IL1RN (P18510) variants and mutations
IL1RN (also known as P18510) is a human protein-coding gene encoding an interleukin-1 receptor antagonist protein. It competitively blocks IL-1 receptor activation without triggering inflammatory signaling, providing an endogenous brake on IL-1-mediated inflammation. Biallelic loss-of-function variants cause deficiency of the IL-1 receptor antagonist, a severe neonatal autoinflammatory disease with skin and bone inflammation. This analysis covers 389 IL1RN variants and mutations. Of these, 95% have computational variant effect predictions. Disease context includes sterile multifocal osteomyelitis with periostitis and pustulosis, gout, and abdominal aortic aneurysm. Example IL1RN variants include M1?, E2K, and p.Glu9del.
Variant analysis overview
- Gene: IL1RN
- Protein: P18510
- UniProt accession: P18510
- Organism: Homo sapiens
- Variants analyzed: 389
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 239 unspecified-consequence records; 73 missense variants; 9 frameshift variants; 58 synonymous variants; 4 in-frame deletions; 2 stop-gained variants; 2 splice-region variants; 2 substitution
- Prediction scores: 368 variants have prediction scores (95% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: sterile multifocal osteomyelitis with periostitis and pustulosis, gout, abdominal aortic aneurysm, diabetic retinopathy, ischemic stroke, coronary artery disorder, venous thromboembolism, autoinflammatory syndrome, hypothyroidism, hypertrophic cardiomyopathy, testicular hydrocele, cervix erosion.
Protein structure and variant hotspots
- Protein features: 1 post-translational modification sites.
- PTM context: 2 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable IL1RN variants
Examples include M1?, E2K, p.Glu9del, E2E, E2V, E2Q, I3F, I3N. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1?, cosmic curated COSV52079
- E2K (p.Glu2Lys), cosmic curated COSV52081, REVEL 0.06, CADD 14.40
- E9del (p.Glu9del), gnomAD 2-113120076-TGAA-, CADD 4.74
- E2E (p.Glu2Glu), gnomAD 2-113120079-A-G, CADD 2.84
- E2V (p.Glu2Val), rs749244809, gnomAD 2-113120081-A-T, MetaLR 0.05, MetaSVM -1.02
- E2Q (p.Glu2Gln), gnomAD 2-113127628-G-C, REVEL 0.05, CADD 14.10
- I3F (p.Ile3Phe), cosmic curated COSV10636, SIFT 0.00
- I3N (p.Ile3Asn), gnomAD 2-113127632-T-A, REVEL 0.05, CADD 9.73
- C4* (p.Cys4Ter), gnomAD 2-113127627-G-GGA, CADD 15.80
- C4R (p.Cys4Arg), gnomAD 2-113127634-T-C, REVEL 0.02, CADD 7.14
- C4F (p.Cys4Phe), gnomAD 2-113127635-G-T, REVEL 0.03, CADD 7.74
- C4C (p.Cys4Cys), gnomAD 2-113127636-C-T, CADD 10.50
- R5T (p.Arg5Thr), cosmic curated COSV10877
- R5* (p.Arg5Ter), gnomAD 2-113127637-A-T, CADD 12.00
- G6C (p.Gly6Cys), cosmic curated COSV99381, SIFT 0.22
- p.Gly14 Gly15del, gnomAD 2-113120082-AGGAG, CADD 5.56
- G6R (p.Gly6Arg), rs770976676, gnomAD 2-113120083-G-C, MetaLR 0.09, MetaSVM -1.00
- G6E (p.Gly6Glu), rs1463856176, gnomAD 2-113120084-G-A, MetaLR 0.09, MetaSVM -1.02
- G6G (p.Gly6Gly), gnomAD 2-113120085-A-G, CADD 6.57
- G6S (p.Gly6Ser), gnomAD 2-113120086-G-A, MetaLR 0.06, MetaSVM -0.98
- G6D (p.Gly6Asp), gnomAD 2-113120087-G-A, MetaLR 0.09, MetaSVM -1.00
- G6A (p.Gly6Ala), rs1284620319, gnomAD 2-113120093-G-C, MetaLR 0.06, MetaSVM -0.96
- G6V (p.Gly6Val), gnomAD 2-113120105-G-T, MetaLR 0.05, MetaSVM -1.03
- L7F (p.Leu7Phe), gnomAD rs1224903381, REVEL 0.02, CADD 2.52
- L7* (p.Leu7Ter), gnomAD 2-113118023-CT-C, CADD 15.80
- L7I (p.Leu7Ile), rs1293345956, gnomAD 2-113118025-T-A, MetaLR 0.05, MetaSVM -1.05
- L7V (p.Leu7Val), gnomAD 2-113118025-T-G, MetaLR 0.05, MetaSVM -1.04
- L7S (p.Leu7Ser), rs1373711868, gnomAD 2-113118026-T-C, MetaLR 0.07, MetaSVM -0.99
- L7L (p.Leu7Leu), gnomAD 2-113120073-G-A, CADD 0.41
- R8C (p.Arg8Cys), cosmic curated COSV52082, ESP rs372736558, ExAC rs372736558, TOPMed rs372736558, REVEL 0.01, CADD 0.12
- R8H (p.Arg8His), rs538999895, ClinGen CA1838741, ClinVar RCV000513390, 1000Genomes rs538999895, REVEL 0.06, CADD 0.43, Likely benign, not provided
- R8L (p.Arg8Leu), 1000Genomes rs538999895, ExAC rs538999895, TOPMed rs538999895, gnomAD rs538999895, REVEL 0.07, CADD 0.34, Likely benign
- R8R (p.Arg8Arg), gnomAD 2-113127648-C-T, CADD 6.95
- S9G (p.Ser9Gly), 1000Genomes rs199841275, ESP rs199841275, ExAC rs199841275, TOPMed rs199841275, REVEL 0.01, CADD 3.28
- S9I (p.Ser9Ile), cosmic curated COSV52080, SIFT 0.11
- S9N (p.Ser9Asn), TOPMed rs1240752552, REVEL 0.07, CADD 10.40
- S9R (p.Ser9Arg), 1000Genomes rs199841275, ESP rs199841275, ExAC rs199841275, TOPMed rs199841275, REVEL 0.01, CADD 2.95
- H10Q (p.His10Gln), TOPMed rs1687008924, SIFT 0.16
- H10H (p.His10His), gnomAD 2-113127654-C-T, CADD 13.80
- L11I (p.Leu11Ile), TOPMed rs1275778229, gnomAD rs1275778229, REVEL 0.26, CADD 10.80
- L11P (p.Leu11Pro), TOPMed rs1483659610, gnomAD rs1483659610, REVEL 0.43, CADD 15.20
- L11V (p.Leu11Val), TOPMed rs1275778229, gnomAD rs1275778229, REVEL 0.28, CADD 11.00
- L11L (p.Leu11Leu), rs1204532963, gnomAD 2-113127657-A-G, CADD 9.01
- I12F (p.Ile12Phe), TOPMed rs1687009513
- I12T (p.Ile12Thr), Ensembl rs1687009647, SIFT 0.01
- I12I (p.Ile12Ile), rs758927925, gnomAD 2-113127660-C-T, CADD 8.00
- T13A (p.Thr13Ala), TOPMed rs1687009924, SIFT 0.20
- T13T (p.Thr13Thr), rs368716176, gnomAD 2-113127663-T-A, CADD 8.27
- L14L (p.Leu14Leu), rs1687010354, gnomAD 2-113127666-C-T, CADD 5.09
- L15F (p.Leu15Phe), gnomAD rs1490908524, REVEL 0.07, CADD 10.20
- L15P (p.Leu15Pro), Ensembl rs1687010626, SIFT 0.00
- L15L (p.Leu15Leu), rs767074604, gnomAD 2-113127669-C-G, CADD 14.30
- L16F (p.Leu16Phe), cosmic curated COSV52079, SIFT 0.15
- L16del (p.Leu16del), rs750031723, gnomAD 2-113127663-TCTC-, CADD 12.00
- L16V (p.Leu16Val), gnomAD 2-113127670-C-G, REVEL 0.07, CADD 14.40
- L16P (p.Leu16Pro), gnomAD 2-113127671-T-C, REVEL 0.26, CADD 17.60
- F17C (p.Phe17Cys), gnomAD 2-113127674-T-G, REVEL 0.22, CADD 17.20
- L18V (p.Leu18Val), ExAC rs752268718, gnomAD rs752268718, REVEL 0.15, CADD 15.40
- L18L (p.Leu18Leu), gnomAD 2-113127676-C-T, CADD 15.60
- L18P (p.Leu18Pro), gnomAD 2-113127677-T-C, REVEL 0.34, CADD 17.00
- F19L (p.Phe19Leu), rs970470359, ClinGen CA53692952, ClinVar RCV003629762, TOPMed rs970470359, REVEL 0.10, CADD 10.40, Likely benign, not specified; Sterile multifocal osteomyelitis with periostitis and pustulosis
- H20Y (p.His20Tyr), cosmic curated COSV52081, ExAC rs755803786, gnomAD rs755803786, REVEL 0.03, CADD 10.90
- S21* (p.Ser21Ter), rs112879651, ClinGen CA53692982, cosmic curated COSV52081, ClinVar RCV000512716, CADD 19.00, Likely pathogenic
- S21L (p.Ser21Leu), cosmic curated COSV10726, REVEL 0.14, CADD 14.70
- S21S (p.Ser21Ser), gnomAD 2-113120124-A-G, CADD 1.86
- E22V (p.Glu22Val), NCI-TCGA TCGA novel, MetaLR 0.14, MetaSVM -0.74, Variant assessed as somatic; moderate impact.
- E22G (p.Glu22Gly), rs1686716995, gnomAD 2-113120102-A-G, MetaLR 0.05, MetaSVM -1.08
- E22D (p.Glu22Asp), gnomAD 2-113120103-A-C, MetaLR 0.04, MetaSVM -1.05
- E22K (p.Glu22Lys), gnomAD 2-113120107-G-A, MetaLR 0.05, MetaSVM -1.02
- E22Q (p.Glu22Gln), rs373740711, gnomAD 2-113120128-G-C, MetaLR 0.08, MetaSVM -1.01
- T23M (p.Thr23Met), rs55860727, ClinGen CA1838751, cosmic curated COSV99381, ClinVar RCV001027789, REVEL 0.17, MetaLR 0.26, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis; Microvascular
- T23T (p.Thr23Thr), gnomAD 2-113127693-G-C, CADD 1.65
- I24M (p.Ile24Met), ExAC rs778651108, TOPMed rs778651108, gnomAD rs778651108, REVEL 0.02, MetaLR 0.05
- I24N (p.Ile24Asn), rs1687011890, ClinGen CA348293634, ClinVar RCV003369793, REVEL 0.02, MetaLR 0.04, Uncertain significance, Inborn genetic diseases
- I24T (p.Ile24Thr), Ensembl rs1687011890, MetaLR 0.04, MetaSVM -1.04
- I24V (p.Ile24Val), Ensembl rs2104451905, REVEL 0.03, MetaLR 0.04
- I24L (p.Ile24Leu), gnomAD 2-113127689-AGACG, CADD 24.40
- I24S (p.Ile24Ser), gnomAD 2-113127692-CG-C, CADD 12.30
- C25Y (p.Cys25Tyr), gnomAD rs1406422984, REVEL 0.12, MetaLR 0.15
- R26* (p.Arg26Ter), ExAC rs745852014, TOPMed rs745852014, gnomAD rs745852014, CADD 34.00
- R26P (p.Arg26Pro), rs758363942, ClinGen CA1838755, ClinVar RCV004405151, ExAC rs758363942, REVEL 0.05, MetaLR 0.06, Uncertain significance, Inborn genetic diseases
- R26Q (p.Arg26Gln), rs758363942, ClinGen CA1838756, NCI-TCGA Cosmic COSV5208, cosmic curated COSV52080, REVEL 0.01, MetaLR 0.06, Uncertain significance, Autoinflammatory syndrome; Inborn genetic diseases; Sterile multifocal osteomyel
- R26R (p.Arg26Arg), rs745852014, gnomAD 2-113127700-C-A, CADD 3.57
- P27A (p.Pro27Ala), ExAC rs747206860, TOPMed rs747206860, gnomAD rs747206860, REVEL 0.13, MetaLR 0.14, Uncertain significance
- P27H (p.Pro27His), ExAC rs777003410, gnomAD rs777003410, REVEL 0.15, MetaLR 0.26
- P27L (p.Pro27Leu), ExAC rs777003410, gnomAD rs777003410, REVEL 0.18, MetaLR 0.25, Uncertain significance, Inborn genetic diseases
- P27S (p.Pro27Ser), rs747206860, ClinGen CA1838757, ClinVar RCV000646721, ClinVar RCV005348171, REVEL 0.10, MetaLR 0.15, Uncertain significance, Inborn genetic diseases; Sterile multifocal osteomyelitis with periostitis and p
- P27P (p.Pro27Pro), gnomAD 2-113127705-C-T, CADD 1.85
- S28C (p.Ser28Cys), ESP rs147288195, ExAC rs147288195, TOPMed rs147288195, gnomAD rs147288195, REVEL 0.01, MetaLR 0.07, Uncertain significance, Inborn genetic diseases
- S28A (p.Ser28Ala), gnomAD 2-113127706-T-G, REVEL 0.03, MetaLR 0.04
- S28P (p.Ser28Pro), gnomAD 2-113127706-T-C, REVEL 0.03, MetaLR 0.07
- S28S (p.Ser28Ser), rs1687012785, gnomAD 2-113127708-T-C, CADD 0.55
- G29E (p.Gly29Glu), 1000Genomes rs553560604, ExAC rs553560604, gnomAD rs553560604, REVEL 0.09, MetaLR 0.11
- G29V (p.Gly29Val), NCI-TCGA TCGA novel, MetaLR 0.07, MetaSVM -1.06, Variant assessed as somatic; moderate impact.
- G29R (p.Gly29Arg), gnomAD 2-113127709-G-A, REVEL 0.05, MetaLR 0.11
- G29G (p.Gly29Gly), rs1222799853, gnomAD 2-113127711-G-A, CADD 2.40
- R30T (p.Arg30Thr), gnomAD rs1687013013, REVEL 0.04, MetaLR 0.05
- K31I (p.Lys31Ile), NCI-TCGA TCGA novel, MetaLR 0.05, MetaSVM -1.07, Variant assessed as somatic; moderate impact.
- K31R (p.Lys31Arg), TOPMed rs1687013104, gnomAD rs1687013104, REVEL 0.06, MetaLR 0.01
- K31E (p.Lys31Glu), rs201759499, gnomAD 2-113120125-A-G, MetaLR 0.05, MetaSVM -1.02
- K31N (p.Lys31Asn), gnomAD 2-113120127-G-T, MetaLR 0.06, MetaSVM -1.03
- S32F (p.Ser32Phe), cosmic curated COSV10438
- S32S (p.Ser32Ser), gnomAD 2-113127720-C-A, CADD 3.82
- S33G (p.Ser33Gly), rs1687013175, ClinGen CA348293724, ClinVar RCV002596723, TOPMed rs1687013175, AlphaMissense 0.06, MetaLR 0.05, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis
- S33R (p.Ser33Arg), rs573468124, ClinGen CA1838762, ClinVar RCV002018397, 1000Genomes rs573468124, REVEL 0.03, MetaLR 0.07, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis
- S33I (p.Ser33Ile), gnomAD 2-113127722-G-T, REVEL 0.01, MetaLR 0.07
- K34R (p.Lys34Arg), gnomAD 2-113127725-A-G, REVEL 0.02, MetaLR 0.05
- M35I (p.Met35Ile), ExAC rs763563701, gnomAD rs763563701
- M35L (p.Met35Leu), NCI-TCGA Cosmic COSV9938, cosmic curated COSV99381, TOPMed rs1361738311, gnomAD rs1361738311, Variant assessed as somatic; moderate impact.
- M35T (p.Met35Thr), cosmic curated COSV52080
- M35V (p.Met35Val), TOPMed rs1361738311, gnomAD rs1361738311, MetaLR 0.10, MetaSVM -0.89
- Q36K (p.Gln36Lys), cosmic curated COSV10726, MetaLR 0.03, MetaSVM -1.02
- Q36P (p.Gln36Pro), Ensembl rs968463490, REVEL 0.07, MetaLR 0.03
- Q36Q (p.Gln36Gln), rs144691672, gnomAD 2-113127732-A-G, CADD 8.53
- A37D (p.Ala37Asp), ExAC rs775132427, gnomAD rs775132427, REVEL 0.13, MetaLR 0.03, Uncertain significance, Inborn genetic diseases
- A37S (p.Ala37Ser), rs1573301763, ClinGen CA348293774, ClinVar RCV000813494, Ensembl rs1573301763, AlphaMissense 0.09, MetaLR 0.03, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis
- A37T (p.Ala37Thr), rs1226009223, gnomAD 2-113118022-G-A, MetaLR 0.08, MetaSVM -1.02
- A37P (p.Ala37Pro), rs1383677539, gnomAD 2-113118028-G-C, MetaLR 0.09, MetaSVM -1.05
- A37V (p.Ala37Val), gnomAD 2-113120117-C-T, MetaLR 0.05, MetaSVM -1.03
- A37G (p.Ala37Gly), rs775797091, gnomAD 2-113120117-C-G, MetaLR 0.05, MetaSVM -1.04
- A37A (p.Ala37Ala), rs201934089, gnomAD 2-113120118-T-C, CADD 0.72
- F38F (p.Phe38Phe), rs139856782, gnomAD 2-113127738-C-T, CADD 22.30
- R39K (p.Arg39Lys), cosmic curated COSV52080, Ensembl rs1687014223, REVEL 0.12, MetaLR 0.06
- I40F (p.Ile40Phe), gnomAD rs1395406278, REVEL 0.21, MetaLR 0.05
- I40I (p.Ile40Ile), gnomAD 2-113129579-C-A, CADD 11.40
- W41* (p.Trp41Ter), cosmic curated COSV10458
- W41C (p.Trp41Cys), Ensembl rs2104455672
- W41L (p.Trp41Leu), cosmic curated COSV52081, MetaLR 0.06, MetaSVM -1.09
- W41R (p.Trp41Arg), TOPMed rs893020323, REVEL 0.15, MetaLR 0.06
- D42A (p.Asp42Ala), TOPMed rs1336529271, gnomAD rs1336529271, REVEL 0.39, MetaLR 0.15
- D42E (p.Asp42Glu), ExAC rs766285518, gnomAD rs766285518, REVEL 0.27, MetaLR 0.13
- D42G (p.Asp42Gly), rs144607130, gnomAD 2-113120111-A-G, MetaLR 0.06, MetaSVM -0.98
- D42D (p.Asp42Asp), gnomAD 2-113120112-C-T, CADD 1.33
- D42Y (p.Asp42Tyr), gnomAD 2-113120119-G-T, MetaLR 0.05, MetaSVM -0.98
- D42N (p.Asp42Asn), gnomAD 2-113120119-G-A, MetaLR 0.05, MetaSVM -1.04
- V43D (p.Val43Asp), ExAC rs755071562, TOPMed rs755071562, gnomAD rs755071562, REVEL 0.28, MetaLR 0.03
- V43G (p.Val43Gly), ExAC rs755071562, TOPMed rs755071562, gnomAD rs755071562, REVEL 0.24, MetaLR 0.04
- V43A (p.Val43Ala), gnomAD 2-113129587-T-C, REVEL 0.13, MetaLR 0.02
- V43V (p.Val43Val), rs781464453, gnomAD 2-113129588-T-C, CADD 6.12
- N44H (p.Asn44His), rs369994270, gnomAD 2-113120113-A-C, MetaLR 0.06, MetaSVM -1.05
- N44S (p.Asn44Ser), rs149439584, gnomAD 2-113120114-A-G, MetaLR 0.04, MetaSVM -1.00
- N44N (p.Asn44Asn), gnomAD 2-113120115-T-C, CADD 2.59
- Q45* (p.Gln45Ter), rs1019766125, ClinGen CA53694871, NCI-TCGA Cosmic COSV5208, cosmic curated COSV52080, CADD 44.00, Pathogenic
- Q45K (p.Gln45Lys), TOPMed rs1019766125, gnomAD rs1019766125, REVEL 0.16, MetaLR 0.06, Pathogenic
- Q45R (p.Gln45Arg), gnomAD 2-113129593-A-G, REVEL 0.20, MetaLR 0.06
- Q45Q (p.Gln45Gln), gnomAD 2-113129594-G-A, CADD 12.20
- K46N (p.Lys46Asn), gnomAD 2-113129597-G-C, REVEL 0.24, MetaLR 0.09
- T47A (p.Thr47Ala), gnomAD 2-113129598-A-G, REVEL 0.11, MetaLR 0.02
- T47T (p.Thr47Thr), rs2104455713, gnomAD 2-113129600-C-G, CADD 9.63
- F48C (p.Phe48Cys), TOPMed rs1687087517, MetaLR 0.08, MetaSVM -1.09
- F48S (p.Phe48Ser), rs1011480433, gnomAD 2-113129598-AC-A, CADD 24.20
- F48L (p.Phe48Leu), gnomAD 2-113129603-C-G, REVEL 0.18, MetaLR 0.02
- Y49C (p.Tyr49Cys), TOPMed rs1687087705, REVEL 0.34, MetaLR 0.09
- Y49H (p.Tyr49His), rs2466954053, ClinGen CA348294472, ClinVar RCV002614523, REVEL 0.29, MetaLR 0.08, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis
- L50M (p.Leu50Met), NCI-TCGA Cosmic COSV9938, cosmic curated COSV99381, MetaLR 0.04, MetaSVM -1.03, Variant assessed as somatic; moderate impact.
- L50R (p.Leu50Arg), gnomAD rs1687087901, REVEL 0.33, MetaLR 0.10
- L50V (p.Leu50Val), gnomAD 2-113129607-C-G, REVEL 0.15, MetaLR 0.03
- L50L (p.Leu50Leu), rs1687087815, gnomAD 2-113129607-C-T, CADD 10.20
- N52K (p.Asn52Lys), TOPMed rs1022748861, gnomAD rs1022748861, REVEL 0.17, MetaLR 0.06, Likely benign
- N52Y (p.Asn52Tyr), TOPMed rs1687088005, gnomAD rs1687088005, REVEL 0.21, MetaLR 0.08
- N52I (p.Asn52Ile), gnomAD 2-113129614-A-T, REVEL 0.19, MetaLR 0.07
- N52N (p.Asn52Asn), rs1022748861, gnomAD 2-113129615-C-T, CADD 6.07
- N53S (p.Asn53Ser), 1000Genomes rs114647664, MetaLR 0.03, MetaSVM -1.03
- N53N (p.Asn53Asn), rs756418307, gnomAD 2-113129618-C-T, CADD 8.52
- Q54* (p.Gln54Ter), rs121913162, ClinGen CA124205, ClinVar RCV000015790, ClinVar RCV000084164, Pathogenic
- Q54N (p.Gln54Asn), gnomAD 2-113129617-AC-A, CADD 23.90
- L55I (p.Leu55Ile), gnomAD rs1289272328, REVEL 0.19, MetaLR 0.15
- L55Q (p.Leu55Gln), gnomAD 2-113129623-T-A, REVEL 0.44, MetaLR 0.17
- V56I (p.Val56Ile), rs557348234, ClinGen CA53694937, ClinVar RCV001132305, 1000Genomes rs557348234, REVEL 0.03, MetaLR 0.02, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis
- V56L (p.Val56Leu), 1000Genomes rs557348234, TOPMed rs557348234, gnomAD rs557348234, REVEL 0.09, MetaLR 0.02, Uncertain significance
- V56A (p.Val56Ala), gnomAD 2-113129626-T-C, REVEL 0.16, MetaLR 0.07
- V56V (p.Val56Val), gnomAD 2-113129627-T-A, CADD 0.11
- A57S (p.Ala57Ser), rs777996358, ClinGen CA1838797, ClinVar RCV001220016, ExAC rs777996358, REVEL 0.24, MetaLR 0.10, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis
- A57T (p.Ala57Thr), gnomAD 2-113129628-G-A, REVEL 0.29, MetaLR 0.10
- A57A (p.Ala57Ala), rs419598, gnomAD 2-113129630-T-C, CADD 2.54
- G58E (p.Gly58Glu), TOPMed rs1281227831, gnomAD rs1281227831, REVEL 0.39, MetaLR 0.09, Uncertain significance
- G58R (p.Gly58Arg), ExAC rs771212516, gnomAD rs771212516, REVEL 0.39, MetaLR 0.09
- G58V (p.Gly58Val), rs1281227831, ClinGen CA348294619, ClinVar RCV001873903, TOPMed rs1281227831, REVEL 0.33, MetaLR 0.07, Uncertain significance, Sterile multifocal osteomyelitis with periostitis and pustulosis
- G58G (p.Gly58Gly), rs779342025, gnomAD 2-113129633-A-T, CADD 1.68
- Y59C (p.Tyr59Cys), TOPMed rs1687089535, MetaLR 0.07, MetaSVM -1.10
Public IL1RN analysis runs
- IL1RN analysis run — IL1RN (389 variants) — completed 2026-08-19