MBP (Myelin basic protein) variants and mutations
MBP (also known as Myelin basic protein) is a human protein-coding gene encoding a myelin basic protein. It compacts the cytoplasmic surfaces of myelin membranes and helps maintain the multilamellar structure required for rapid nerve conduction. Immune responses against myelin basic protein have long been studied in demyelinating disease, although common human multiple sclerosis is not caused by MBP mutations. This analysis covers 689 MBP variants and mutations. Of these, 80% have computational variant effect predictions. Disease context includes alcohol drinking, duodenal ulcer, and device complication. Example MBP variants include G2R, N3K, and N3T.
Variant analysis overview
- Gene: MBP
- Protein: Myelin basic protein
- UniProt accession: P02686
- Organism: Homo sapiens
- Variants analyzed: 689
- Variant scope: all variants
- Completed: 2026-08-22
Variant and mutation evidence
- Variant composition: 408 unspecified-consequence records; 1 stop retained variant; 171 missense variants; 66 synonymous variants; 23 frameshift variants; 5 in-frame deletions; 5 stop-gained variants; 3 splice-region variants; 3 stop lost; 2 in-frame insertions; 6 substitution
- Prediction scores: 552 variants have prediction scores (80% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: alcohol drinking, duodenal ulcer, device complication, Abnormality of the dentition, preeclampsia, Hepatitis, placenta praevia, pericarditis, myeloid sarcoma, Alzheimer disease, chronic myelogenous leukemia, BCR-ABL1 positive, systemic lupus erythematosus.
Protein structure and variant hotspots
- Protein features: 39 post-translational modification sites.
- PTM context: 94 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable MBP variants
Examples include G2R, N3K, N3T, H4Y, A5G, A5S, A5T, G6S. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- G2R (p.Gly2Arg), cosmic curated COSV10467
- N3K (p.Asn3Lys), Ensembl rs868131695
- N3T (p.Asn3Thr), Ensembl rs1976227731
- H4Y (p.His4Tyr), TOPMed rs947135999, REVEL 0.16, CADD 23.60
- A5G (p.Ala5Gly), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A5S (p.Ala5Ser), 1000Genomes rs149191307, ESP rs149191307, ExAC rs149191307, TOPMed rs149191307, REVEL 0.05, CADD 7.45
- A5T (p.Ala5Thr), cosmic curated COSV63558, 1000Genomes rs149191307, ESP rs149191307, ExAC rs149191307, REVEL 0.04, CADD 9.18
- G6S (p.Gly6Ser), cosmic curated COSV63557
- R8* (p.Arg8Ter), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10059, CADD 35.00, Variant assessed as somatic; high impact.
- R8L (p.Arg8Leu), cosmic curated COSV63559, REVEL 0.22, CADD 25.20
- R8Q (p.Arg8Gln), cosmic curated COSV63556, ExAC rs200267661, TOPMed rs200267661, gnomAD rs200267661, REVEL 0.13, CADD 23.80
- R8R (p.Arg8Arg), rs929755123, []
- E9* (p.Glu9Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- L10* (p.Leu10Ter), cosmic curated COSV63559
- N11D (p.Asn11Asp), TOPMed rs1976226589
- N11K (p.Asn11Lys), NCI-TCGA TCGA novel, REVEL 0.01, CADD 0.00, Variant assessed as somatic; moderate impact.
- A12S (p.Ala12Ser), cosmic curated COSV63559
- A12V (p.Ala12Val), rs747162845, NCI-TCGA Cosmic COSV6355, cosmic curated COSV63557, ExAC rs747162845, REVEL 0.09, CADD 9.87, Variant assessed as somatic; moderate impact.
- E13* (p.Glu13Ter), cosmic curated COSV63556, ExAC rs779270491, TOPMed rs779270491, gnomAD rs779270491, CADD 35.00
- E13K (p.Glu13Lys), ExAC rs779270491, TOPMed rs779270491, gnomAD rs779270491, REVEL 0.11, CADD 18.70
- E13Q (p.Glu13Gln), ExAC rs779270491, TOPMed rs779270491, gnomAD rs779270491, REVEL 0.04, CADD 14.10
- K14E (p.Lys14Glu), TOPMed rs973802590, REVEL 0.11, CADD 22.60
- K14T (p.Lys14Thr), TOPMed rs959367050, REVEL 0.14, CADD 22.50
- A15D (p.Ala15Asp), ExAC rs750008587, gnomAD rs750008587, REVEL 0.03, CADD 8.37
- A15T (p.Ala15Thr), Ensembl rs202054986, REVEL 0.07, CADD 5.48
- S16G (p.Ser16Gly), TOPMed rs1599254873, REVEL 0.12, CADD 7.06
- S16R (p.Ser16Arg), TOPMed rs1976225414
- T17K (p.Thr17Lys), 1000Genomes rs143996211, ESP rs143996211, ExAC rs143996211, TOPMed rs143996211, REVEL 0.10, CADD 14.60
- T17M (p.Thr17Met), 1000Genomes rs143996211, ESP rs143996211, ExAC rs143996211, TOPMed rs143996211, REVEL 0.06, CADD 21.80
- N18D (p.Asn18Asp), gnomAD rs1167148076, REVEL 0.03, CADD 3.68
- N18S (p.Asn18Ser), ExAC rs768186985, TOPMed rs768186985, gnomAD rs768186985, REVEL 0.05, CADD 4.80
- S19R (p.Ser19Arg), Ensembl rs1974200282
- T21A (p.Thr21Ala), ExAC rs748802759, gnomAD rs748802759, REVEL 0.07, CADD 0.01
- N22K (p.Asn22Lys), cosmic curated COSV63559
- R23G (p.Arg23Gly), TOPMed rs1408415487, REVEL 0.03, CADD 10.60
- G24E (p.Gly24Glu), TOPMed rs1401525409, gnomAD rs1401525409, REVEL 0.25, CADD 17.10
- E25* (p.Glu25Ter), cosmic curated COSV10442
- E25K (p.Glu25Lys), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10059, NCI-TCGA Cosmic COSV1044, Variant assessed as somatic; moderate impact.
- S26P (p.Ser26Pro), ExAC rs780036086, TOPMed rs780036086, gnomAD rs780036086, REVEL 0.04, CADD 1.41
- K28N (p.Lys28Asn), cosmic curated COSV63558
- K29N (p.Lys29Asn), cosmic curated COSV10059, TOPMed rs1456775504, gnomAD rs1456775504
- K29R (p.Lys29Arg), TOPMed rs1974199234
- R30K (p.Arg30Lys), gnomAD rs1974199149
- N31K (p.Asn31Lys), 1000Genomes rs1974199060, gnomAD rs1974199060, cosmic curated COSV63556, REVEL 0.02, CADD 6.11
- L35F (p.Leu35Phe), ExAC rs780985755, TOPMed rs780985755, gnomAD rs780985755, REVEL 0.08, CADD 12.80
- S36* (p.Ser36Ter), TOPMed rs1434389370
- S36P (p.Ser36Pro), TOPMed rs1283234002, gnomAD rs1283234002, REVEL 0.11, CADD 5.38
- R37L (p.Arg37Leu), ESP rs145675270, ExAC rs145675270, TOPMed rs145675270, gnomAD rs145675270
- R37P (p.Arg37Pro), ESP rs145675270, ExAC rs145675270, TOPMed rs145675270, gnomAD rs145675270, REVEL 0.17, CADD 0.16
- R37Q (p.Arg37Gln), ESP rs145675270, ExAC rs145675270, TOPMed rs145675270, gnomAD rs145675270, REVEL 0.04, CADD 0.01
- R37W (p.Arg37Trp), rs1242231426, NCI-TCGA Cosmic COSV6355, cosmic curated COSV63559, TOPMed rs1242231426, REVEL 0.14, CADD 21.40, Variant assessed as somatic; moderate impact.
- R37H (p.Arg37His), rs747036508, gnomAD 18-76984796-C-T, CADD 7.43
- R37C (p.Arg37Cys), rs944959302, []
- T38K (p.Thr38Lys), TOPMed rs1974198041
- S40N (p.Ser40Asn), rs572017418, gnomAD 18-76984778-C-T, CADD 2.94
- E41K (p.Glu41Lys), ExAC rs758491700, gnomAD rs758491700, REVEL 0.16, CADD 20.20
- E41V (p.Glu41Val), NCI-TCGA Cosmic COSV6355, cosmic curated COSV63556, Variant assessed as somatic; moderate impact.
- N43K (p.Asn43Lys), ExAC rs760137415, TOPMed rs760137415, gnomAD rs760137415, REVEL 0.08, CADD 2.97
- N43S (p.Asn43Ser), ExAC rs752790125, TOPMed rs752790125, gnomAD rs752790125, REVEL 0.05, CADD 0.10
- E44K (p.Glu44Lys), TOPMed rs1599173711, gnomAD rs1599173711, REVEL 0.14, CADD 16.90
- E44Q (p.Glu44Gln), TOPMed rs1599173711, gnomAD rs1599173711
- E44G (p.Glu44Gly), gnomAD 18-76980463-T-C, CADD 16.90
- E44D (p.Glu44Asp), rs1599445391, gnomAD 18-76980465-T-G, CADD 8.36
- V45E (p.Val45Glu), Ensembl rs1042808324
- F46=, rs377221551, NCI-TCGA Cosmic COSV1005, AlphaMissense 0.97, MetaLR 0.21, Variant assessed as somatic; low impact.
- F46L (p.Phe46Leu), cosmic curated COSV10059, ESP rs377221551, ExAC rs377221551, TOPMed rs377221551, REVEL 0.24, CADD 17.60
- G47* (p.Gly47Ter), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10059, NCI-TCGA Cosmic COSV6355, Variant assessed as somatic; high impact.
- G47R (p.Gly47Arg), rs535536627, NCI-TCGA Cosmic COSV1005, NCI-TCGA Cosmic COSV6355, cosmic curated COSV63556, REVEL 0.22, CADD 25.70, Variant assessed as somatic; moderate impact.
- E48D (p.Glu48Asp), ExAC rs763253942, TOPMed rs763253942, gnomAD rs763253942, REVEL 0.09, CADD 23.50
- E48Q (p.Glu48Gln), ExAC rs777446235, gnomAD rs777446235, REVEL 0.11, CADD 24.00
- A49T (p.Ala49Thr), NCI-TCGA Cosmic COSV6282, cosmic curated COSV62829, REVEL 0.19, CADD 22.70, Variant assessed as somatic; moderate impact.
- A49V (p.Ala49Val), rs761965498, gnomAD 18-76980454-G-A, CADD 6.00
- D50G (p.Asp50Gly), TOPMed rs1398322293, gnomAD rs1398322293, REVEL 0.39, CADD 28.20
- A51E (p.Ala51Glu), gnomAD rs1377507467, REVEL 0.33, CADD 21.60
- A51T (p.Ala51Thr), NCI-TCGA TCGA novel, gnomAD rs1971702821, REVEL 0.09, CADD 22.40, Variant assessed as somatic; moderate impact.
- A51V (p.Ala51Val), gnomAD rs1377507467, REVEL 0.13, CADD 13.10
- N52S (p.Asn52Ser), ExAC rs779241556, REVEL 0.16, CADD 7.43
- Q53H (p.Gln53His), ExAC rs755092177, TOPMed rs755092177, gnomAD rs755092177, REVEL 0.20, CADD 21.70
- Q53K (p.Gln53Lys), cosmic curated COSV10059
- Q53R (p.Gln53Arg), TOPMed rs1971701972
- N54K (p.Asn54Lys), ExAC rs754034418, TOPMed rs754034418, gnomAD rs754034418, REVEL 0.19, CADD 25.60
- N55K (p.Asn55Lys), ExAC rs780636959, gnomAD rs780636959
- N55N (p.Asn55Asn), rs1969114824, gnomAD 18-76980423-G-A, CADD 4.68
- G56R (p.Gly56Arg), TOPMed rs934575568, gnomAD rs934575568, REVEL 0.19, CADD 25.20
- G56* (p.Gly56Ter), gnomAD 18-76980410-C-A, CADD 0.05
- G56G (p.Gly56Gly), gnomAD 18-76980414-A-G, CADD 0.26
- G56S (p.Gly56Ser), rs1490958412, gnomAD 18-76980416-C-T, CADD 1.48
- S58F (p.Ser58Phe), cosmic curated COSV62828, 1000Genomes rs140157048, ESP rs140157048, ExAC rs140157048, REVEL 0.18, CADD 23.20
- S59P (p.Ser59Pro), TOPMed rs1487064616, gnomAD rs1487064616, REVEL 0.13, CADD 21.90
- S59S (p.Ser59Ser), gnomAD 18-76980411-G-T, CADD 3.07
- S59A (p.Ser59Ala), rs918346290, []
- Q60* (p.Gln60Ter), NCI-TCGA Cosmic COSV6282, cosmic curated COSV62829, Variant assessed as somatic; high impact.
- D61G (p.Asp61Gly), Ensembl rs909457101, REVEL 0.05, CADD 15.90
- A63V (p.Ala63Val), 1000Genomes rs61742941, ESP rs61742941, ExAC rs61742941, TOPMed rs61742941, REVEL 0.25, CADD 21.20
- V64A (p.Val64Ala), gnomAD 18-76979991-A-G, CADD 6.24
- V64F (p.Val64Phe), gnomAD 18-76979992-C-A, CADD 9.00
- T65A (p.Thr65Ala), gnomAD rs1276378671, REVEL 0.19, CADD 25.10
- S67F (p.Ser67Phe), ExAC rs776127568, gnomAD rs776127568, REVEL 0.40, CADD 27.20
- S67Y (p.Ser67Tyr), ExAC rs776127568, gnomAD rs776127568, REVEL 0.24, CADD 26.20
- S67S (p.Ser67Ser), rs1969111707, gnomAD 18-76980390-A-G, CADD 8.15
- S67Q (p.Ser67Gln), gnomAD 18-76980397-GA-G, CADD 3.16
- S67P (p.Ser67Pro), gnomAD 18-76980398-A-G, CADD 6.57
- S67T (p.Ser67Thr), rs1350908542, gnomAD 18-76980401-A-T, CADD 1.57
- K68N (p.Lys68Asn), gnomAD rs1216909565, REVEL 0.04, CADD 22.80
- K68Q (p.Lys68Gln), ExAC rs770801249, TOPMed rs770801249, gnomAD rs770801249, REVEL 0.06, CADD 23.00
- K68T (p.Lys68Thr), cosmic curated COSV62830
- R69C (p.Arg69Cys), rs1403050775, NCI-TCGA Cosmic COSV6282, cosmic curated COSV62829, TOPMed rs1403050775, REVEL 0.15, CADD 23.70, Variant assessed as somatic; moderate impact.
- R69H (p.Arg69His), rs529411261, NCI-TCGA Cosmic COSV6283, cosmic curated COSV62830, 1000Genomes rs529411261, REVEL 0.05, CADD 16.80, Variant assessed as somatic; moderate impact.
- R69L (p.Arg69Leu), 1000Genomes rs529411261, ExAC rs529411261, TOPMed rs529411261, gnomAD rs529411261, REVEL 0.06, CADD 20.80
- T70A (p.Thr70Ala), cosmic curated COSV62829
- T70T (p.Thr70Thr), gnomAD 18-76980011-C-A, CADD 0.52
- T70M (p.Thr70Met), rs1969089291, gnomAD 18-76980012-G-A, CADD 6.67
- T70K (p.Thr70Lys), gnomAD 18-76980033-G-T, CADD 7.66
- A71E (p.Ala71Glu), ExAC rs748030999, TOPMed rs748030999, gnomAD rs748030999, REVEL 0.03, CADD 7.71
- A71V (p.Ala71Val), rs748030999, NCI-TCGA Cosmic COSV1005, cosmic curated COSV10059, ExAC rs748030999, REVEL 0.14, CADD 10.80, Variant assessed as somatic; moderate impact.
- D72E (p.Asp72Glu), TOPMed rs1971697584
- P73L (p.Pro73Leu), 1000Genomes rs139814021, ESP rs139814021, ExAC rs139814021, TOPMed rs139814021, REVEL 0.40, CADD 25.80
- P73Q (p.Pro73Gln), 1000Genomes rs139814021, ESP rs139814021, ExAC rs139814021, TOPMed rs139814021
- P73R (p.Pro73Arg), 1000Genomes rs139814021, ESP rs139814021, ExAC rs139814021, TOPMed rs139814021, REVEL 0.45, CADD 25.40
- P73S (p.Pro73Ser), TOPMed rs1971697484
- P73T (p.Pro73Thr), rs1969114491, gnomAD 18-76980419-G-T, CADD 0.62
- P73P (p.Pro73Pro), gnomAD 18-76980420-T-C, CADD 0.05
- P73H (p.Pro73His), gnomAD 18-76980420-TG-T, CADD 0.01
- K74M (p.Lys74Met), cosmic curated COSV62828
- K74N (p.Lys74Asn), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10059, REVEL 0.02, CADD 23.20, Variant assessed as somatic; moderate impact.
- K74T (p.Lys74Thr), gnomAD rs1971697032, REVEL 0.15, CADD 23.40
- K74K (p.Lys74Lys), gnomAD 18-76980038-C-T, CADD 2.16
- N75D (p.Asn75Asp), ExAC rs746329133, gnomAD rs746329133, REVEL 0.16, CADD 23.30
- A76G (p.Ala76Gly), Ensembl rs1971696733
- A76T (p.Ala76Thr), Ensembl rs1971696834
- p.Trp86 Thr91del, rs1464744850, gnomAD 18-76979993-AGTCC, CADD 10.50
- W77* (p.Trp77Ter), rs1479671372, gnomAD 18-76980008-C-T, CADD 5.83
- W77L (p.Trp77Leu), rs1310155270, gnomAD 18-76980009-C-A, CADD 5.26
- W77R (p.Trp77Arg), rs1209144688, gnomAD 18-76980010-A-T, CADD 0.08
- W77C (p.Trp77Cys), gnomAD 18-76988294-C-A, CADD 0.29
- Q78H (p.Gln78His), gnomAD rs1169288186, REVEL 0.19, CADD 9.56
- Q78Q (p.Gln78Gln), rs1428393296, gnomAD 18-76979981-T-C, CADD 0.12
- Q78E (p.Gln78Glu), gnomAD 18-76979983-G-C, CADD 9.17
- D79G (p.Asp79Gly), gnomAD rs1971696362, REVEL 0.13, CADD 13.00
- D79V (p.Asp79Val), gnomAD rs1971696362, REVEL 0.12, CADD 14.20
- D79Y (p.Asp79Tyr), TOPMed rs1476565648, gnomAD rs1476565648, REVEL 0.14, CADD 22.90
- A80S (p.Ala80Ser), cosmic curated COSV62830, REVEL 0.38, CADD 22.70
- A80T (p.Ala80Thr), Ensembl rs1971696261, REVEL 0.23, CADD 24.30
- A80V (p.Ala80Val), cosmic curated COSV62829, Ensembl rs868032492, REVEL 0.27, CADD 26.90
- A80A (p.Ala80Ala), gnomAD 18-76980026-T-A, CADD 7.36
- A80D (p.Ala80Asp), rs1485831853, gnomAD 18-76980030-G-T, CADD 7.17
- H81N (p.His81Asn), ExAC rs781748075, gnomAD rs781748075, REVEL 0.07, CADD 13.20
- H81Q (p.His81Gln), 1000Genomes rs150638800, ESP rs150638800, ExAC rs150638800, TOPMed rs150638800, REVEL 0.09, CADD 22.90, Likely benign
- H81H (p.His81His), gnomAD 18-76980035-G-A, CADD 6.80
- P82Q (p.Pro82Gln), cosmic curated COSV10059, REVEL 0.26, CADD 25.90
- A83G (p.Ala83Gly), Ensembl rs866895503, REVEL 0.21, CADD 26.20
- A83T (p.Ala83Thr), rs746208269, gnomAD 18-76980004-C-T, CADD 2.66
- A83S (p.Ala83Ser), gnomAD 18-76980004-C-A, CADD 2.12
- A83A (p.Ala83Ala), rs779654409, gnomAD 18-76980005-C-T, CADD 2.10
- A83E (p.Ala83Glu), gnomAD 18-76980006-G-T, CADD 0.14
- A83V (p.Ala83Val), rs746809343, gnomAD 18-76980006-G-A, CADD 0.22
- D84N (p.Asp84Asn), ExAC rs764803706, TOPMed rs764803706, gnomAD rs764803706, REVEL 0.19, CADD 26.80
- P85L (p.Pro85Leu), cosmic curated COSV10467, REVEL 0.12, CADD 25.10
- P85S (p.Pro85Ser), TOPMed rs1971695481, REVEL 0.04, CADD 21.20
- G86R (p.Gly86Arg), ExAC rs754642326, gnomAD rs754642326, REVEL 0.16, CADD 14.30
- R88C (p.Arg88Cys), rs1206368278, NCI-TCGA Cosmic COSV6282, TOPMed rs1206368278, gnomAD rs1206368278, REVEL 0.46, CADD 32.00, Variant assessed as somatic; moderate impact.
- R88H (p.Arg88His), rs141290653, cosmic curated COSV62828, ESP rs141290653, ExAC rs141290653, REVEL 0.34, CADD 27.20, Variant assessed as somatic; moderate impact.
- R88S (p.Arg88Ser), NCI-TCGA Cosmic COSV6282, cosmic curated COSV62829, Variant assessed as somatic; moderate impact.
- R88D (p.Arg88Asp), rs1969087699, gnomAD 18-76979996-CCT-C, CADD 7.18
- P89A (p.Pro89Ala), ExAC rs765907364, TOPMed rs765907364, gnomAD rs765907364, REVEL 0.50, CADD 25.40
- H90N (p.His90Asn), ExAC rs773007424, gnomAD rs773007424, REVEL 0.51, CADD 25.80
- H90P (p.His90Pro), gnomAD rs1007140529, REVEL 0.29, CADD 26.30
- H90R (p.His90Arg), gnomAD rs1007140529, REVEL 0.30, CADD 25.00
- H90Y (p.His90Tyr), ExAC rs773007424, gnomAD rs773007424, REVEL 0.75, CADD 26.00
- L91L (p.Leu91Leu), gnomAD 18-76980402-C-T, CADD 5.56
- L91P (p.Leu91Pro), rs2123027271, gnomAD 18-76980403-A-G, CADD 0.49
- I92M (p.Ile92Met), gnomAD rs1228024634, REVEL 0.12, CADD 25.10
- I92I (p.Ile92Ile), rs558508660, gnomAD 18-76979984-G-A, CADD 11.50
- I92F (p.Ile92Phe), gnomAD 18-76979986-T-A, CADD 8.37
- I92S (p.Ile92Ser), gnomAD 18-76980406-A-C, CADD 0.35
- I92V (p.Ile92Val), gnomAD 18-76980407-T-C, CADD 2.66
- I92T (p.Ile92Thr), gnomAD 18-76980460-A-G, CADD 7.19
- R93C (p.Arg93Cys), cosmic curated COSV62829, ExAC rs767554831, TOPMed rs767554831, gnomAD rs767554831, REVEL 0.81, CADD 32.00
- R93H (p.Arg93His), ExAC rs761443800, TOPMed rs761443800, gnomAD rs761443800, REVEL 0.55, CADD 28.10
- R93P (p.Arg93Pro), ExAC rs761443800, TOPMed rs761443800, gnomAD rs761443800
Public MBP analysis runs
- MBP analysis run — MBP (689 variants) — completed 2026-08-22