ADCY5 (Adenylate cyclase type 5) variants and mutations
ADCY5 (also known as Adenylate cyclase type 5) is a human protein-coding gene encoding an adenylate cyclase type 5 protein. It generates cyclic AMP downstream of G-protein-coupled receptors and is particularly important in striatal and cardiac signaling. Gain-of-function and loss-of-function variants can both cause movement disorders, with ADCY5-related dyskinesia often featuring episodic chorea, dystonia, and nocturnal exacerbations. This analysis covers 1,842 ADCY5 variants and mutations. Of these, 87% have computational variant effect predictions. Disease context includes dyskinesia with orofacial involvement, autosomal dominant, Familial dyskinesia and facial myokymia, and dyskinesia with orofacial involvement, autosomal recessive. Example ADCY5 variants include G3C, G3S, and S4C.
Variant analysis overview
- Gene: ADCY5
- Protein: Adenylate cyclase type 5
- UniProt accession: O95622
- Organism: Homo sapiens
- Variants analyzed: 1842
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 1,627 unspecified-consequence records; 117 synonymous variants; 79 missense variants; 10 frameshift variants; 4 in-frame deletions; 3 splice-region variants; 1 in-frame insertions; 1 stop-gained variants
- Prediction scores: 1,602 variants have prediction scores (87% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: dyskinesia with orofacial involvement, autosomal dominant, Familial dyskinesia and facial myokymia, dyskinesia with orofacial involvement, autosomal recessive, neurodevelopmental disorder with hyperkinetic movements and dyskinesia, hereditary disease, type 2 diabetes mellitus, diabetes mellitus, dyskinesia with orofacial involvement, chronic obstructive pulmonary disease, diabetic neuropathy, diabetic retinopathy, Dystonia.
Protein structure and variant hotspots
- Protein features: 12 transmembrane segments; 2 domains; 12 binding sites; 8 post-translational modification sites.
- Structural context: 692 variants have structural context.
- PTM context: 14 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable ADCY5 variants
Examples include G3C, G3S, S4C, S4Y, K5N, S6G, S6I, S6N. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- G3C (p.Gly3Cys), TOPMed rs1279127415, gnomAD rs1279127415, REVEL 0.21, MetaLR 0.20, Uncertain significance
- G3S (p.Gly3Ser), rs1279127415, ClinGen CA354359114, ClinVar RCV002676253, TOPMed rs1279127415, REVEL 0.26, MetaLR 0.14, Uncertain significance, not provided
- S4C (p.Ser4Cys), TOPMed rs1945873673, gnomAD rs1945873673, REVEL 0.39, MetaLR 0.43
- S4Y (p.Ser4Tyr), TOPMed rs1945873673, gnomAD rs1945873673, REVEL 0.40, MetaLR 0.41
- K5N (p.Lys5Asn), TOPMed rs1945873630, MetaLR 0.21, MetaSVM -0.93
- S6G (p.Ser6Gly), rs1460670980, ClinGen CA354359093, ClinVar RCV003284973, ClinVar RCV003779917, REVEL 0.26, MetaLR 0.30, Uncertain significance, Inborn genetic diseases; not provided
- S6I (p.Ser6Ile), rs977612868, ClinGen CA82636619, ClinVar RCV001891496, TOPMed rs977612868, REVEL 0.44, MetaLR 0.39, Benign, not provided
- S6N (p.Ser6Asn), rs977612868, ClinGen CA82636622, ClinVar RCV003227362, ClinVar RCV005812113, REVEL 0.36, MetaLR 0.36, Uncertain significance, Inborn genetic diseases; not provided
- S6R (p.Ser6Arg), TOPMed rs1474680093, REVEL 0.27, MetaLR 0.34
- V7L (p.Val7Leu), rs1945873464, ClinGen CA354359086, ClinVar RCV003323120, ClinVar RCV005399327, REVEL 0.27, MetaLR 0.29, Uncertain significance, not provided; Dyskinesia with orofacial involvement, autosomal dominant; Dyskine
- S8I (p.Ser8Ile), rs1945873405, ClinGen CA354359077, ClinVar RCV003118946, ClinVar RCV005554912, REVEL 0.38, MetaLR 0.32, Uncertain significance, not provided; Inborn genetic diseases
- P9A (p.Pro9Ala), rs1382254140, ClinGen CA354359073, ClinVar RCV003019727, REVEL 0.29, MetaLR 0.40, Uncertain significance, not provided
- P9L (p.Pro9Leu), TOPMed rs1945873324, REVEL 0.36, MetaLR 0.42
- P9S (p.Pro9Ser), gnomAD rs1382254140, REVEL 0.29, MetaLR 0.40
- P10L (p.Pro10Leu), rs143905423, ClinGen CA2577748, ClinVar RCV001521983, ClinVar RCV002253837, REVEL 0.43, MetaLR 0.46, Benign/Likely benign, Dyskinesia with orofacial involvement, autosomal recessive; Neurodevelopmental d
- P10R (p.Pro10Arg), 1000Genomes rs143905423, ESP rs143905423, ExAC rs143905423, TOPMed rs143905423, REVEL 0.51, MetaLR 0.58, Benign
- P10S (p.Pro10Ser), TOPMed rs1426562302, REVEL 0.43, MetaLR 0.40, Uncertain significance, Inborn genetic diseases
- Y12H (p.Tyr12His), rs1020556677, ClinGen CA82636582, ClinVar RCV001955538, ClinVar RCV004975954, REVEL 0.23, MetaLR 0.21, Conflicting interpretations, Inborn genetic diseases; not provided
- A13E (p.Ala13Glu), TOPMed rs1324485629, gnomAD rs1324485629, REVEL 0.19, MetaLR 0.22
- A13V (p.Ala13Val), TOPMed rs1324485629, gnomAD rs1324485629, REVEL 0.18, MetaLR 0.22
- A14T (p.Ala14Thr), Ensembl rs1945872873, REVEL 0.20, MetaLR 0.29
- Q15H (p.Gln15His), gnomAD rs1245151733, REVEL 0.27, MetaLR 0.31
- Q15R (p.Gln15Arg), rs1406512689, ClinGen CA354359034, ClinVar RCV002695282, ClinVar RCV004973563, REVEL 0.21, MetaLR 0.19, Conflicting interpretations, not provided; Inborn genetic diseases
- T17A (p.Thr17Ala), Ensembl rs1285607274, REVEL 0.12, MetaLR 0.12
- A18E (p.Ala18Glu), gnomAD rs1945872457, REVEL 0.21, MetaLR 0.19
- A18T (p.Ala18Thr), gnomAD rs1945872536, REVEL 0.23, MetaLR 0.21
- A18V (p.Ala18Val), NCI-TCGA TCGA novel, gnomAD rs1945872457, REVEL 0.16, MetaLR 0.19, Variant assessed as somatic; moderate impact.
- A19T (p.Ala19Thr), rs550254165, ClinGen CA2577747, ClinVar RCV000871723, ClinVar RCV004540235, REVEL 0.19, MetaLR 0.23, Conflicting interpretations, not provided
- A21T (p.Ala21Thr), TOPMed rs1945872220, gnomAD rs1945872220, REVEL 0.20, MetaLR 0.19
- P22S (p.Pro22Ser), TOPMed rs1945872086, REVEL 0.14, MetaLR 0.16
- R23G (p.Arg23Gly), rs1209746484, ClinGen CA354358987, ClinVar RCV002788193, ClinVar RCV003777751, REVEL 0.13, MetaLR 0.21, Conflicting interpretations, not provided; Inborn genetic diseases
- R23W (p.Arg23Trp), 1000Genomes rs1209746484, TOPMed rs1209746484, gnomAD rs1209746484, REVEL 0.30, MetaLR 0.25, Benign
- G24A (p.Gly24Ala), TOPMed rs939696995, MetaLR 0.22, MetaSVM -0.81
- P26L (p.Pro26Leu), rs752897516, ClinGen CA2577746, ClinVar RCV001879559, ExAC rs752897516, REVEL 0.21, MetaLR 0.22, Conflicting interpretations, not provided
- P26R (p.Pro26Arg), ExAC rs752897516, TOPMed rs752897516, gnomAD rs752897516, REVEL 0.21, MetaLR 0.22, Uncertain significance
- H28Q (p.His28Gln), rs1007815586, TOPMed rs1007815586, gnomAD rs1007815586, ClinGen CA354358952, REVEL 0.28, MetaLR 0.20, Uncertain significance, not provided
- R29H (p.Arg29His), TOPMed rs1945871408, REVEL 0.32, MetaLR 0.43
- R29L (p.Arg29Leu), TOPMed rs1945871408, REVEL 0.36, MetaLR 0.35
- S30F (p.Ser30Phe), rs1455983225, ClinGen CA354358940, ClinVar RCV003156649, TOPMed rs1455983225, REVEL 0.34, MetaLR 0.34, Uncertain significance, not provided
- A31V (p.Ala31Val), gnomAD rs1945871343, REVEL 0.25, MetaLR 0.35
- E34Q (p.Glu34Gln), rs1559883468, ClinGen CA354358917, ClinVar RCV000714656, Ensembl rs1559883468, AlphaMissense 0.19, MetaLR 0.42, Uncertain significance, Dyskinesia with orofacial involvement, autosomal dominant
- E34V (p.Glu34Val), TOPMed rs1332675880, gnomAD rs1332675880, REVEL 0.39, MetaLR 0.34
- D36H (p.Asp36His), ExAC rs779142923, TOPMed rs779142923, gnomAD rs779142923, REVEL 0.23, MetaLR 0.23, Uncertain significance
- D36N (p.Asp36Asn), ExAC rs779142923, TOPMed rs779142923, gnomAD rs779142923, REVEL 0.27, MetaLR 0.20, Uncertain significance, Dyskinesia with orofacial involvement, autosomal dominant
- D36Y (p.Asp36Tyr), ExAC rs779142923, TOPMed rs779142923, gnomAD rs779142923, REVEL 0.30, MetaLR 0.23, Uncertain significance
- S37A (p.Ser37Ala), TOPMed rs908234617, gnomAD rs908234617, REVEL 0.17, MetaLR 0.23
- S37C (p.Ser37Cys), TOPMed rs1945871079, REVEL 0.41, MetaLR 0.31
- R38C (p.Arg38Cys), TOPMed rs1945871038, REVEL 0.28, MetaLR 0.24
- R38H (p.Arg38His), gnomAD rs1394490827, REVEL 0.31, MetaLR 0.27
- N40H (p.Asn40His), TOPMed rs1945870941, gnomAD rs1945870941, REVEL 0.29, MetaLR 0.35
- N40K (p.Asn40Lys), Ensembl rs1576705041, REVEL 0.25, MetaLR 0.28
- N40S (p.Asn40Ser), gnomAD rs1167400845, REVEL 0.32, MetaLR 0.29
- Y42* (p.Tyr42Ter), gnomAD rs1161865354, CADD 36.00
- Y42C (p.Tyr42Cys), TOPMed rs1370443253, gnomAD rs1370443253, REVEL 0.18, MetaLR 0.16
- Y42N (p.Tyr42Asn), TOPMed rs1945870813, gnomAD rs1945870813, REVEL 0.24, MetaLR 0.23
- Y42S (p.Tyr42Ser), TOPMed rs1370443253, gnomAD rs1370443253, REVEL 0.23, MetaLR 0.22
- P43L (p.Pro43Leu), gnomAD rs1443826183, REVEL 0.26, MetaLR 0.24
- H44N (p.His44Asn), rs189868197, ClinGen CA2577744, ClinVar RCV003732130, 1000Genomes rs189868197, REVEL 0.21, MetaLR 0.14, Likely benign, not provided
- H44Y (p.His44Tyr), rs189868197, ClinGen CA2577743, ClinVar RCV000870961, ClinVar RCV002507514, REVEL 0.13, MetaLR 0.04, Benign/Likely benign, Dyskinesia with orofacial involvement, autosomal recessive; Neurodevelopmental d
- A45D (p.Ala45Asp), ExAC rs761040973, REVEL 0.19, MetaLR 0.20
- A45S (p.Ala45Ser), ExAC rs766890471, gnomAD rs766890471, REVEL 0.13, MetaLR 0.13, Uncertain significance
- A45T (p.Ala45Thr), rs766890471, ClinGen CA354358846, ClinVar RCV001884707, ExAC rs766890471, REVEL 0.17, MetaLR 0.18, Uncertain significance, not provided
- P46L (p.Pro46Leu), TOPMed rs1357790160, gnomAD rs1357790160, REVEL 0.23, MetaLR 0.22
- G47A (p.Gly47Ala), rs1945870281, ClinGen CA354358833, ClinVar RCV004371165, REVEL 0.11, MetaLR 0.14, Uncertain significance, Inborn genetic diseases
- G47E (p.Gly47Glu), gnomAD rs1945870281, REVEL 0.16, MetaLR 0.15, Uncertain significance, Inborn genetic diseases
- G47R (p.Gly47Arg), 1000Genomes rs564518568, TOPMed rs564518568, REVEL 0.16, MetaLR 0.13
- G47W (p.Gly47Trp), 1000Genomes rs564518568, TOPMed rs564518568, REVEL 0.33, MetaLR 0.21, Uncertain significance, not provided
- G48D (p.Gly48Asp), TOPMed rs1310429137, gnomAD rs1310429137, REVEL 0.32, MetaLR 0.16
- G48S (p.Gly48Ser), ExAC rs750822850, gnomAD rs750822850, REVEL 0.24, MetaLR 0.14
- G48V (p.Gly48Val), TOPMed rs1310429137, gnomAD rs1310429137, REVEL 0.28, MetaLR 0.22
- S49A (p.Ser49Ala), rs921195392, ClinGen CA82636455, ClinVar RCV002120207, ClinVar RCV003025420, REVEL 0.11, MetaLR 0.22, Conflicting interpretations, not provided; Inborn genetic diseases
- S49F (p.Ser49Phe), rs762609054, ClinGen CA2577737, ClinVar RCV001913610, ClinVar RCV004042838, REVEL 0.27, MetaLR 0.25, Conflicting interpretations, Inborn genetic diseases; not provided; not specified
- A50T (p.Ala50Thr), ExAC rs775111352, gnomAD rs775111352, REVEL 0.19, MetaLR 0.15
- A50V (p.Ala50Val), TOPMed rs1328717130, gnomAD rs1328717130, REVEL 0.19, MetaLR 0.20
- R51C (p.Arg51Cys), TOPMed rs975210243, gnomAD rs975210243, REVEL 0.32, MetaLR 0.31
- R51H (p.Arg51His), TOPMed rs1301581448, gnomAD rs1301581448, REVEL 0.33, MetaLR 0.29
- R51S (p.Arg51Ser), TOPMed rs975210243, gnomAD rs975210243, REVEL 0.30, MetaLR 0.27
- G52D (p.Gly52Asp), gnomAD rs1380755130, REVEL 0.16, MetaLR 0.23
- G52R (p.Gly52Arg), TOPMed rs1945869596, REVEL 0.15, MetaLR 0.20
- G52S (p.Gly52Ser), TOPMed rs1945869596, Uncertain significance, Inborn genetic diseases
- S53F (p.Ser53Phe), gnomAD rs1468357680, REVEL 0.26, MetaLR 0.24
- S53P (p.Ser53Pro), Ensembl rs1945869481, REVEL 0.16, MetaLR 0.21
- T54A (p.Thr54Ala), rs2473329745, ClinGen CA354358799, ClinVar RCV002949005, REVEL 0.14, MetaLR 0.14, Uncertain significance, not provided
- K55E (p.Lys55Glu), gnomAD rs1292378035, REVEL 0.23, MetaLR 0.23
- K55N (p.Lys55Asn), TOPMed rs968289964, gnomAD rs968289964, REVEL 0.27, MetaLR 0.23
- P57S (p.Pro57Ser), rs1199435756, ClinGen CA354358777, ClinVar RCV002015660, TOPMed rs1199435756, REVEL 0.14, MetaLR 0.11, Uncertain significance, not provided
- G58A (p.Gly58Ala), ExAC rs769256576, gnomAD rs769256576, REVEL 0.08, MetaLR 0.19
- G59E (p.Gly59Glu), Ensembl rs2107659284, REVEL 0.07, MetaLR 0.15
- G59R (p.Gly59Arg), rs1184128181, ClinGen CA354358768, ClinVar RCV002246943, 1000Genomes rs1184128181, REVEL 0.16, MetaLR 0.18, Uncertain significance, not specified
- A60G (p.Ala60Gly), TOPMed rs1022376951, gnomAD rs1022376951, REVEL 0.15, MetaLR 0.21
- A60S (p.Ala60Ser), gnomAD rs1221350025, REVEL 0.15, MetaLR 0.16
- A60V (p.Ala60Val), NCI-TCGA TCGA novel, TOPMed rs1022376951, gnomAD rs1022376951, REVEL 0.14, MetaLR 0.22, Variant assessed as somatic; moderate impact.
- V61L (p.Val61Leu), NCI-TCGA TCGA novel, REVEL 0.11, MetaLR 0.18, Variant assessed as somatic; moderate impact.
- T62I (p.Thr62Ile), Ensembl rs1945868860, REVEL 0.36, MetaLR 0.31
- T62P (p.Thr62Pro), Ensembl rs1559883333, REVEL 0.35, MetaLR 0.21
- P63A (p.Pro63Ala), ExAC rs759057691, gnomAD rs759057691, REVEL 0.28, MetaLR 0.33
- P63L (p.Pro63Leu), TOPMed rs1415710264, gnomAD rs1415710264, REVEL 0.36, MetaLR 0.34
- Q64P (p.Gln64Pro), rs1010098398, ClinGen CA16604438, ClinVar RCV000435389, ClinVar RCV005318388, REVEL 0.24, MetaLR 0.16, Uncertain significance, Inborn genetic diseases; not provided
- Q64S (p.Gln64Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- Q65R (p.Gln65Arg), TOPMed rs956718156, REVEL 0.17, MetaLR 0.17
- Q66H (p.Gln66His), TOPMed rs1945868597, REVEL 0.11, MetaLR 0.18
- Q66P (p.Gln66Pro), TOPMed rs1945868637, REVEL 0.28, MetaLR 0.18, Uncertain significance, not provided
- R68G (p.Arg68Gly), gnomAD rs1348937614, REVEL 0.39, MetaLR 0.30, Likely pathogenic, not provided
- R68H (p.Arg68His), rs776480737, ClinGen CA354358707, ClinVar RCV002030944, ExAC rs776480737, REVEL 0.23, MetaLR 0.29, Uncertain significance, not provided
- R68L (p.Arg68Leu), ExAC rs776480737, TOPMed rs776480737, gnomAD rs776480737, REVEL 0.35, MetaLR 0.27, Uncertain significance
- R68P (p.Arg68Pro), rs776480737, ClinGen CA2577731, ClinVar RCV001794739, ExAC rs776480737, REVEL 0.28, MetaLR 0.28, Conflicting interpretations, not provided
- L69V (p.Leu69Val), gnomAD rs1343489621
- A70P (p.Ala70Pro), rs559947047, ClinGen CA2577727, ClinVar RCV001787494, 1000Genomes rs559947047, REVEL 0.24, MetaLR 0.25, Conflicting interpretations, not provided
- A70S (p.Ala70Ser), 1000Genomes rs559947047, ExAC rs559947047, TOPMed rs559947047, gnomAD rs559947047, REVEL 0.21, MetaLR 0.18, Uncertain significance
- A70T (p.Ala70Thr), 1000Genomes rs559947047, ExAC rs559947047, TOPMed rs559947047, gnomAD rs559947047, REVEL 0.20, MetaLR 0.24, Uncertain significance
- A70V (p.Ala70Val), gnomAD rs1945868086, REVEL 0.19, MetaLR 0.22
- S71R (p.Ser71Arg), ExAC rs777714893, TOPMed rs777714893, gnomAD rs777714893, REVEL 0.12, MetaLR 0.28, Likely benign
- R72G (p.Arg72Gly), gnomAD rs1281450842, REVEL 0.34, MetaLR 0.28
- R72H (p.Arg72His), ExAC rs771931187, TOPMed rs771931187, gnomAD rs771931187, REVEL 0.38, MetaLR 0.37, Uncertain significance, not provided
- R72L (p.Arg72Leu), rs771931187, ClinGen CA2577725, ClinVar RCV003836670, ClinVar RCV004366872, REVEL 0.24, MetaLR 0.30, Uncertain significance, Inborn genetic diseases; not provided
- W73* (p.Trp73Ter), gnomAD rs1300219097, CADD 36.00
- W73C (p.Trp73Cys), NCI-TCGA TCGA novel, REVEL 0.48, MetaLR 0.43, Variant assessed as somatic; moderate impact.
- W73G (p.Trp73Gly), ExAC rs779269584, TOPMed rs779269584, gnomAD rs779269584, REVEL 0.44, MetaLR 0.32
- W73R (p.Trp73Arg), ExAC rs779269584, TOPMed rs779269584, gnomAD rs779269584, REVEL 0.47, MetaLR 0.37
- R74C (p.Arg74Cys), NCI-TCGA TCGA novel, REVEL 0.57, MetaLR 0.47, Uncertain significance, not provided
- R74G (p.Arg74Gly), Ensembl rs1945867668
- R74L (p.Arg74Leu), ExAC rs755064886, gnomAD rs755064886, REVEL 0.47, MetaLR 0.43
- S75R (p.Ser75Arg), TOPMed rs1945867505, gnomAD rs1945867505, REVEL 0.13, MetaLR 0.20
- S75T (p.Ser75Thr), gnomAD rs1383929179, REVEL 0.11, MetaLR 0.18
- D76H (p.Asp76His), rs753975649, ClinGen CA2577721, ClinVar RCV002856871, ClinVar RCV004064967, REVEL 0.25, MetaLR 0.34, Conflicting interpretations, Inborn genetic diseases; not provided
- D77V (p.Asp77Val), rs1945867183, ClinGen CA354358652, ClinVar RCV001320429, Ensembl rs1945867183, REVEL 0.19, MetaLR 0.29, Uncertain significance, not provided
- D78G (p.Asp78Gly), rs1477827448, ClinGen CA354358644, ClinVar RCV002621404, TOPMed rs1477827448, REVEL 0.23, MetaLR 0.30, Likely benign, not provided
- D78N (p.Asp78Asn), ExAC rs756652189, gnomAD rs756652189, REVEL 0.20, MetaLR 0.32
- D78Y (p.Asp78Tyr), ExAC rs756652189, gnomAD rs756652189, REVEL 0.35, MetaLR 0.41
- D79E (p.Asp79Glu), ESP rs371231929, TOPMed rs371231929, gnomAD rs371231929, REVEL 0.17, MetaLR 0.14
- D79G (p.Asp79Gly), NCI-TCGA TCGA novel, REVEL 0.18, MetaLR 0.19, Variant assessed as somatic; moderate impact.
- D79N (p.Asp79Asn), gnomAD rs1264925299, REVEL 0.17, MetaLR 0.15
- D79Y (p.Asp79Tyr), gnomAD rs1264925299, REVEL 0.17, MetaLR 0.16
- D80G (p.Asp80Gly), gnomAD rs1186182344, REVEL 0.26, MetaLR 0.23
- D80H (p.Asp80His), rs750872257, ClinGen CA354358633, ClinVar RCV003739625, ExAC rs750872257, REVEL 0.27, MetaLR 0.24, Uncertain significance, not provided
- D80N (p.Asp80Asn), ExAC rs750872257, TOPMed rs750872257, gnomAD rs750872257, REVEL 0.20, MetaLR 0.22, Uncertain significance
- D80V (p.Asp80Val), gnomAD rs1186182344, REVEL 0.29, MetaLR 0.23
- D80Y (p.Asp80Tyr), ExAC rs750872257, TOPMed rs750872257, gnomAD rs750872257, REVEL 0.26, MetaLR 0.23, Uncertain significance
- P81L (p.Pro81Leu), rs77439349, ClinGen CA2577716, ClinVar RCV001513381, ClinVar RCV002295342, REVEL 0.14, MetaLR 0.21, Conflicting interpretations, Dyskinesia with orofacial involvement, autosomal dominant; Dyskinesia with orofa
- P82L (p.Pro82Leu), ExAC rs762162693, TOPMed rs762162693, gnomAD rs762162693, REVEL 0.17, MetaLR 0.21
- P82Q (p.Pro82Gln), ExAC rs762162693, TOPMed rs762162693, gnomAD rs762162693, REVEL 0.22, MetaLR 0.20
- P82S (p.Pro82Ser), TOPMed rs1261754830, gnomAD rs1261754830, REVEL 0.24, MetaLR 0.19
- P82T (p.Pro82Thr), rs1261754830, ClinGen CA354358621, ClinVar RCV002592806, REVEL 0.26, MetaLR 0.17, Uncertain significance, not provided
- G85R (p.Gly85Arg), rs764919392, ClinGen CA354358599, ClinVar RCV003328804, ExAC rs764919392, REVEL 0.25, MetaLR 0.18, Uncertain significance, not provided
- G85S (p.Gly85Ser), ExAC rs764919392, TOPMed rs764919392, gnomAD rs764919392, REVEL 0.19, MetaLR 0.19, Uncertain significance
- D86V (p.Asp86Val), Ensembl rs1945866450, REVEL 0.16, MetaLR 0.16
- D87Y (p.Asp87Tyr), rs529481040, ClinGen CA2577712, ClinVar RCV001950272, ClinVar RCV004043082, REVEL 0.14, MetaLR 0.20, Conflicting interpretations, not provided; Inborn genetic diseases
- P88L (p.Pro88Leu), NCI-TCGA Cosmic COSV1015, Ensembl rs1945866257, REVEL 0.21, MetaLR 0.26, Uncertain significance, not provided
- P88S (p.Pro88Ser), gnomAD rs1415889532, REVEL 0.15, MetaLR 0.16, Uncertain significance, Inborn genetic diseases
- L89V (p.Leu89Val), ExAC rs770280288, gnomAD rs770280288, REVEL 0.12, MetaLR 0.16
- A90T (p.Ala90Thr), ExAC rs773265276, gnomAD rs773265276, REVEL 0.12, MetaLR 0.15, Uncertain significance, Inborn genetic diseases
- A90V (p.Ala90Val), TOPMed rs1338819669, gnomAD rs1338819669, REVEL 0.17, MetaLR 0.15
- G91R (p.Gly91Arg), ExAC rs772055808, TOPMed rs772055808, gnomAD rs772055808, REVEL 0.19, MetaLR 0.22
- G92D (p.Gly92Asp), TOPMed rs1485287534, gnomAD rs1485287534, REVEL 0.10, MetaLR 0.20
- G92V (p.Gly92Val), TOPMed rs1485287534, gnomAD rs1485287534, REVEL 0.04, MetaLR 0.14
- S96R (p.Ser96Arg), ExAC rs773970900, gnomAD rs773970900, REVEL 0.24, MetaLR 0.33
- S96T (p.Ser96Thr), TOPMed rs899367992, REVEL 0.21, MetaLR 0.35, Uncertain significance, not provided
- R98C (p.Arg98Cys), ExAC rs749408400, TOPMed rs749408400, gnomAD rs749408400, REVEL 0.63, MetaLR 0.36
- R98S (p.Arg98Ser), ExAC rs749408400, TOPMed rs749408400, gnomAD rs749408400, REVEL 0.39, MetaLR 0.31
- K100E (p.Lys100Glu), ExAC rs780200428, TOPMed rs780200428, gnomAD rs780200428, REVEL 0.41, MetaLR 0.29
- K100M (p.Lys100Met), TOPMed rs1038111568, gnomAD rs1038111568, REVEL 0.36, MetaLR 0.30, Uncertain significance
- K100N (p.Lys100Asn), ExAC rs756174070, TOPMed rs756174070, gnomAD rs756174070, REVEL 0.27, MetaLR 0.29
- K100Q (p.Lys100Gln), ExAC rs780200428, TOPMed rs780200428, gnomAD rs780200428, REVEL 0.39, MetaLR 0.30
- K100T (p.Lys100Thr), rs1038111568, ClinGen CA82636278, ClinVar RCV001587694, TOPMed rs1038111568, REVEL 0.45, MetaLR 0.32, Uncertain significance, not provided
- S101F (p.Ser101Phe), TOPMed rs1190923336, gnomAD rs1190923336, REVEL 0.34, MetaLR 0.31
- A102S (p.Ala102Ser), 1000Genomes rs548282891, ExAC rs548282891, TOPMed rs548282891, gnomAD rs548282891, REVEL 0.20, MetaLR 0.29, Benign
- A102T (p.Ala102Thr), rs548282891, ClinGen CA2577700, ClinVar RCV000428751, ClinVar RCV000765702, REVEL 0.21, MetaLR 0.28, Conflicting interpretations, Inborn genetic diseases; not provided; Dyskinesia with orofacial involvement, au
- W103* (p.Trp103Ter), TOPMed rs1945865120, CADD 37.00, Uncertain significance
- W103L (p.Trp103Leu), rs1945865120, ClinGen CA354358403, ClinVar RCV003698314, TOPMed rs1945865120, REVEL 0.47, MetaLR 0.41, Uncertain significance, not provided
- W103R (p.Trp103Arg), gnomAD rs1338982718, REVEL 0.33, MetaLR 0.41
- Q104K (p.Gln104Lys), gnomAD rs1284940679, REVEL 0.19, MetaLR 0.31
- Q104L (p.Gln104Leu), ExAC rs781642194, TOPMed rs781642194, gnomAD rs781642194, REVEL 0.23, MetaLR 0.30
- Q104R (p.Gln104Arg), ExAC rs781642194, TOPMed rs781642194, gnomAD rs781642194, REVEL 0.14, MetaLR 0.30, Uncertain significance, not provided
- R106C (p.Arg106Cys), rs2107659076, ClinGen CA354358371, ClinVar RCV001774476, NCI-TCGA TCGA novel, REVEL 0.29, MetaLR 0.19, Uncertain significance, not provided
- R106P (p.Arg106Pro), ExAC rs757669816, gnomAD rs757669816, REVEL 0.14, MetaLR 0.18
- G107A (p.Gly107Ala), gnomAD rs1447414292, REVEL 0.09, MetaLR 0.25
- G107R (p.Gly107Arg), ExAC rs751941964, gnomAD rs751941964, REVEL 0.09, MetaLR 0.25
- G107V (p.Gly107Val), rs1447414292, ClinGen CA354358358, ClinVar RCV003578427, REVEL 0.14, MetaLR 0.28, Uncertain significance, not provided
- D109E (p.Asp109Glu), rs868724293, ClinGen CA82636265, ClinVar RCV003388806, gnomAD rs868724293, REVEL 0.09, MetaLR 0.10, Uncertain significance, not provided
- D109G (p.Asp109Gly), rs1373192640, ClinGen CA354358339, ClinVar RCV002730680, REVEL 0.13, MetaLR 0.21, Uncertain significance, not provided
Public ADCY5 analysis runs
- ADCY5 analysis run — ADCY5 (1,842 variants) — completed 2026-08-19