RIT1 (GTP-binding protein Rit1) variants and mutations
RIT1 (also known as GTP-binding protein Rit1) is a human protein-coding gene encoding a GTP-binding protein. It transmits growth and stress signals through RAS-MAPK and related pathways and is important in cardiovascular and nervous-system development. Germline activating variants cause Noonan syndrome, often with a high frequency of hypertrophic cardiomyopathy. This analysis covers 534 RIT1 variants and mutations. Of these, 88% have computational variant effect predictions. Disease context includes Noonan syndrome, RASopathy, and Noonan syndrome and Noonan-related syndrome. Example RIT1 variants include M1?, D2A, and D2E.
Variant analysis overview
- Gene: RIT1
- Protein: GTP-binding protein Rit1
- UniProt accession: Q92963
- Organism: Homo sapiens
- Variants analyzed: 534
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 334 unspecified-consequence records; 1 stop retained variant; 82 synonymous variants; 91 missense variants; 10 frameshift variants; 4 in-frame deletions; 2 stop-gained variants; 5 splice-region variants; 5 substitution
- Prediction scores: 469 variants have prediction scores (88% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Noonan syndrome, RASopathy, Noonan syndrome and Noonan-related syndrome, Abnormality of the cardiovascular system, hereditary disease, Non-immune hydrops fetalis, congenital heart disease, Short stature, Pedal edema, Hypertelorism, Downslanted palpebral fissures, megalencephaly-capillary malformation-polymicrogyria syndrome.
Protein structure and variant hotspots
- Protein features: 15 binding sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable RIT1 variants
Examples include M1?, D2A, D2E, D2G, D2N, S3A, S3F, G4A. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1?, NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- D2A (p.Asp2Ala), Ensembl rs1673578900
- D2E (p.Asp2Glu), TOPMed rs1673578848
- D2G (p.Asp2Gly), cosmic curated COSV10085, SIFT 0.41
- D2N (p.Asp2Asn), rs924364497, ClinGen CA30950977, ClinVar RCV001879186, TOPMed rs924364497, REVEL 0.11, CADD 20.30, Uncertain significance, Noonan syndrome 8
- S3A (p.Ser3Ala), rs2102591265, ClinGen CA342776577, ClinVar RCV002034404, Ensembl rs2102591265, AlphaMissense 0.06, MetaLR 0.04, Uncertain significance, Noonan syndrome 8
- S3F (p.Ser3Phe), ExAC rs775310783, gnomAD rs775310783, REVEL 0.11, CADD 19.40
- G4A (p.Gly4Ala), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G4E (p.Gly4Glu), rs2102591253, ClinGen CA342776563, ClinVar RCV001932288, ClinVar RCV004656689, REVEL 0.26, CADD 19.40, Uncertain significance, Noonan syndrome 8; Cardiovascular phenotype
- G4R (p.Gly4Arg), rs2102591257, ClinGen CA342776568, ClinVar RCV001937057, ClinVar RCV006280837, AlphaMissense 0.18, MetaLR 0.07, Uncertain significance, not provided; Noonan syndrome 8
- T5I (p.Thr5Ile), rs2527198125, ClinGen CA342776545, ClinVar RCV003741821, Uncertain significance, Noonan syndrome 8
- T5S (p.Thr5Ser), rs771768320, ClinGen CA1151911, ClinVar RCV000820043, ClinVar RCV002390686, REVEL 0.05, CADD 0.04, Uncertain significance, Cardiovascular phenotype; Noonan syndrome 8
- R6G (p.Arg6Gly), Ensembl rs1373221300
- R6H (p.Arg6His), TOPMed rs1255067143, gnomAD rs1255067143, REVEL 0.21, CADD 22.90, Uncertain significance
- R6P (p.Arg6Pro), rs1255067143, ClinGen CA342776536, ClinVar RCV002586590, TOPMed rs1255067143, REVEL 0.24, CADD 23.00, Uncertain significance, Noonan syndrome 8
- p.Arg6 Val8del, rs1673578086, gnomAD 1-155910737-CAACT, CADD 16.40
- R6R (p.Arg6Arg), rs1376159930, gnomAD 1-155910744-G-A, CADD 9.92
- P7L (p.Pro7Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P7Q (p.Pro7Gln), cosmic curated COSV10592
- P7S (p.Pro7Ser), NCI-TCGA TCGA novel, SIFT 0.06, Variant assessed as somatic; moderate impact.
- V8A (p.Val8Ala), rs977203137, ClinGen CA342776508, ClinVar RCV003740770, ClinVar RCV003909118, REVEL 0.04, CADD 0.15, Uncertain significance, Noonan syndrome 8
- V8F (p.Val8Phe), rs1193358245, ClinGen CA342776512, ClinVar RCV002446313, ClinVar RCV003741315, REVEL 0.16, CADD 9.72, Uncertain significance, Noonan syndrome 8; Cardiovascular phenotype
- V8G (p.Val8Gly), TOPMed rs977203137, Uncertain significance, Noonan syndrome 8
- V8I (p.Val8Ile), gnomAD rs1193358245, REVEL 0.13, CADD 9.78, Uncertain significance, not provided
- V8L (p.Val8Leu), cosmic curated COSV10468
- G9G (p.Gly9Gly), gnomAD 1-155910735-A-G, CADD 3.70
- G9R (p.Gly9Arg), gnomAD 1-155910737-C-G, REVEL 0.14, CADD 19.90
- G9S (p.Gly9Ser), gnomAD 1-155910737-C-T, REVEL 0.14, CADD 19.40
- S10I (p.Ser10Ile), rs1673577896, ClinGen CA342776484, ClinVar RCV002282884, AlphaMissense 0.12, MetaLR 0.12, Uncertain significance, not specified
- S10N (p.Ser10Asn), Ensembl rs1673577896, REVEL 0.19, AlphaMissense 0.12
- S10G (p.Ser10Gly), ExAC rs745465435, gnomAD rs745465435, REVEL 0.08, CADD 9.02, Uncertain significance, Cardiovascular phenotype
- S10R (p.Ser10Arg), cosmic curated COSV64167
- S10T (p.Ser10Thr), rs1673577896, ClinGen CA342776485, ClinVar RCV003847127, AlphaMissense 0.12, MetaLR 0.12, Uncertain significance, Noonan syndrome 8
- S10S (p.Ser10Ser), gnomAD 1-155910732-G-A, CADD 13.10
- S10L (p.Ser10Leu), rs1673578024, gnomAD 1-155910733-CTA-C, CADD 17.10
- C11* (p.Cys11Ter), cosmic curated COSV10970
- C11C (p.Cys11Cys), rs968579100, gnomAD 1-155910729-G-A, CADD 9.53
- C12G (p.Cys12Gly), ExAC rs773931858, gnomAD rs773931858, REVEL 0.04, CADD 12.40
- C12S (p.Cys12Ser), rs1177306699, ClinGen CA342776449, ClinVar RCV004079516, REVEL 0.09, CADD 9.81, Uncertain significance, Cardiovascular phenotype
- C12Y (p.Cys12Tyr), rs1177306699, ClinGen CA342776452, ClinVar RCV001905488, ClinVar RCV005472951, REVEL 0.08, CADD 15.30, Conflicting interpretations, Cardiovascular phenotype; Noonan syndrome 8
- S13N (p.Ser13Asn), rs145034964, ClinGen CA1151908, ClinVar RCV001697491, ClinVar RCV001813519, REVEL 0.04, CADD 17.60, Conflicting interpretations, Noonan syndrome and Noonan-related syndrome; Cardiovascular phenotype; Noonan sy
- S13R (p.Ser13Arg), cosmic curated COSV64167, REVEL 0.08, CADD 18.90
- S14I (p.Ser14Ile), rs1673577435, ClinGen CA342776413, ClinVar RCV002327859, REVEL 0.07, CADD 20.30, Uncertain significance, Cardiovascular phenotype
- S14N (p.Ser14Asn), rs1673577435, ClinGen CA342776417, ClinVar RCV002327856, TOPMed rs1673577435, REVEL 0.10, CADD 14.50, Uncertain significance, Cardiovascular phenotype
- P15L (p.Pro15Leu), gnomAD rs1271650033, REVEL 0.09, CADD 21.20
- P15P (p.Pro15Pro), rs748838734, gnomAD 1-155910717-G-C, CADD 5.02
- P15R (p.Pro15Arg), gnomAD 1-155910718-G-C, REVEL 0.07, CADD 17.50
- A16T (p.Ala16Thr), rs1131692009, ClinGen CA342776396, ClinVar RCV000494418, ClinVar RCV002329177, REVEL 0.05, CADD 13.40, Uncertain significance, Cardiovascular phenotype; not provided; Noonan syndrome 8
- A16S (p.Ala16Ser), gnomAD 1-155910716-C-A, REVEL 0.03, CADD 8.51
- G17E (p.Gly17Glu), rs2527197964, ClinGen CA342776381, ClinVar RCV003741897, Uncertain significance, Noonan syndrome 8
- G17W (p.Gly17Trp), cosmic curated COSV10468, Uncertain significance, Noonan syndrome 8
- G17G (p.Gly17Gly), rs1346635558, gnomAD 1-155910711-C-T, CADD 9.26
- L18H (p.Leu18His), gnomAD 1-155910709-A-T, REVEL 0.11, CADD 19.40
- L18F (p.Leu18Phe), gnomAD 1-155910710-G-A, REVEL 0.12, CADD 18.80
- S19* (p.Ser19Ter), cosmic curated COSV64167
- S19L (p.Ser19Leu), NCI-TCGA Cosmic COSV6416, cosmic curated COSV64167, SIFT 0.87, Variant assessed as somatic; moderate impact.
- S19T (p.Ser19Thr), rs1277754109, gnomAD 1-155910705-TGA-T, CADD 27.30
- R20Q (p.Arg20Gln), cosmic curated COSV64167, ExAC rs778233462, gnomAD rs778233462, SIFT 0.02, Uncertain significance, Noonan syndrome 8
- R20W (p.Arg20Trp), gnomAD rs1409117266, REVEL 0.46, CADD 24.20, Uncertain significance, Cardiovascular phenotype
- R20R (p.Arg20Arg), gnomAD 1-155910702-C-T, CADD 8.64
- E21D (p.Glu21Asp), TOPMed rs1571999532, SIFT 0.21
- E21S (p.Glu21Ser), rs747459574, gnomAD 1-155910700-TC-T, CADD 26.90
- Y22D (p.Tyr22Asp), Ensembl rs1571999524, Uncertain significance, not provided
- K23E (p.Lys23Glu), rs869312687, ClinGen CA342776314, NCI-TCGA Cosmic COSV6416, cosmic curated COSV64166, AlphaMissense 0.99, MetaLR 0.73, Pathogenic, Noonan syndrome 8
- K23N (p.Lys23Asn), rs1557962794, ClinGen CA342776306, ClinVar RCV000704832, ClinVar RCV000856799, AlphaMissense 0.99, MetaLR 0.56, Pathogenic, Noonan syndrome 8; Noonan syndrome 1; not provided
- K23Q (p.Lys23Gln), rs869312687, ClinGen CA353413, ClinVar RCV000209835, ClinVar RCV000521893, AlphaMissense 0.99, MetaLR 0.73, Pathogenic/Likely pathogenic, Cardiovascular phenotype; Hypertelorism; Short stature
- K23R (p.Lys23Arg), gnomAD rs1311275491, REVEL 0.71, CADD 25.20
- L24L (p.Leu24Leu), rs770237120, gnomAD 1-155910690-T-C, CADD 7.71
- L24V (p.Leu24Val), gnomAD 1-155910692-G-C, REVEL 0.33, CADD 17.60
- V25V (p.Val25Val), gnomAD 1-155910687-C-T, CADD 16.10
- M26I (p.Met26Ile), rs2527197889, ClinGen CA342776271, ClinVar RCV003236569, Uncertain significance, not specified
- A29S (p.Ala29Ser), cosmic curated COSV64166, SIFT 0.54
- A29T (p.Ala29Thr), gnomAD 1-155910677-C-T, REVEL 0.28, CADD 23.70
- G30V (p.Gly30Val), cosmic curated COSV64167, REVEL 0.52, CADD 25.10
- G30A (p.Gly30Ala), gnomAD 1-155910673-C-G, REVEL 0.44, CADD 24.70
- G30D (p.Gly30Asp), gnomAD 1-155910673-C-T, REVEL 0.54, CADD 25.10
- G31R (p.Gly31Arg), rs1571999498, ClinGen CA342776221, ClinVar RCV000856810, ClinVar RCV003396492, REVEL 0.66, CADD 25.40, Pathogenic/Likely pathogenic, Noonan syndrome 1; Noonan syndrome 8; RIT1-related disorder
- G31V (p.Gly31Val), TOPMed rs1673576237, REVEL 0.72, CADD 24.80
- G31A (p.Gly31Ala), gnomAD 1-155910670-C-G, REVEL 0.60, CADD 24.30
- G31C (p.Gly31Cys), gnomAD 1-155910671-C-A, REVEL 0.67, CADD 26.00
- V32I (p.Val32Ile), gnomAD 1-155910668-C-T, REVEL 0.53, CADD 24.00
- G33G (p.Gly33Gly), rs199914900, gnomAD 1-155910663-C-T, CADD 5.51
- K34M (p.Lys34Met), NCI-TCGA Cosmic COSV6416, Variant assessed as somatic; moderate impact.
- K34N (p.Lys34Asn), NCI-TCGA Cosmic COSV6416, cosmic curated COSV64166, Variant assessed as somatic; moderate impact.
- K34T (p.Lys34Thr), cosmic curated COSV64166, SIFT 0.02
- S35T (p.Ser35Thr), rs869025189, ClinGen CA353872, ClinVar RCV000207341, ClinVar RCV000255076, REVEL 0.59, CADD 24.00, Pathogenic, Noonan syndrome; RASopathy; Noonan syndrome 8
- S35S (p.Ser35Ser), rs1335151363, gnomAD 1-155910657-A-G, CADD 1.77
- A36=, NCI-TCGA Cosmic COSV1008, Variant assessed as somatic; low impact.
- A36G (p.Ala36Gly), TOPMed rs1490178310, gnomAD rs1490178310, REVEL 0.86, CADD 32.00
- A36V (p.Ala36Val), cosmic curated COSV10943
- A36A (p.Ala36Ala), rs962881455, gnomAD 1-155910505-G-A, CADD 17.50
- M37V (p.Met37Val), Ensembl rs1557962700, SIFT 1.00, Uncertain significance, Noonan syndrome 8
- T38A (p.Thr38Ala), rs1557962699, ClinGen CA342776100, NCI-TCGA Cosmic COSV6416, cosmic curated COSV64167, AlphaMissense 0.86, MetaLR 0.39, Conflicting interpretations, not specified; not provided; Noonan syndrome 8
- T38I (p.Thr38Ile), rs2102590960, ClinGen CA342776096, ClinVar RCV002451793, AlphaMissense 0.93, MetaLR 0.45, Uncertain significance, Cardiovascular phenotype
- T38N (p.Thr38Asn), rs2102590960, ClinGen CA342776093, ClinVar RCV001261139, ClinVar RCV002541575, AlphaMissense 0.93, MetaLR 0.45, Conflicting interpretations, Noonan syndrome 8
- T38S (p.Thr38Ser), rs2102590960, ClinGen CA342776094, ClinVar RCV001362346, ClinVar RCV001732138, REVEL 0.76, AlphaMissense 0.93, Conflicting interpretations, Noonan syndrome 8; not specified
- M39I (p.Met39Ile), rs748634085, ClinGen CA1151882, ClinVar RCV004517221, ExAC rs748634085, REVEL 0.45, CADD 21.70, Uncertain significance, Cardiovascular phenotype
- M39K (p.Met39Lys), rs2102590945, ClinGen CA342776084, cosmic curated COSV10943, ClinVar RCV001373704, AlphaMissense 0.97, MetaLR 0.30, Uncertain significance, Noonan syndrome 8
- M39R (p.Met39Arg), rs2102590945, ClinGen CA342776082, ClinVar RCV001730034, Ensembl rs2102590945, AlphaMissense 0.97, MetaLR 0.30, Conflicting interpretations, Noonan syndrome 8
- M39T (p.Met39Thr), rs2102590945, ClinGen CA342776085, ClinVar RCV001807974, ClinVar RCV004040927, REVEL 0.70, AlphaMissense 0.97, Uncertain significance, Cardiovascular phenotype; Noonan syndrome 8
- M39V (p.Met39Val), rs769298435, ClinGen CA1151883, ClinVar RCV002373186, ExAC rs769298435, REVEL 0.36, CADD 22.10, Uncertain significance, Cardiovascular phenotype
- Q40* (p.Gln40Ter), rs1057518189, ClinGen CA16042341, ClinVar RCV000414539, Ensembl rs1057518189, Uncertain significance
- Q40L (p.Gln40Leu), cosmic curated COSV64166, SIFT 0.00
- Q40Q (p.Gln40Gln), rs1015730634, gnomAD 1-155910493-C-T, CADD 13.10
- F41L (p.Phe41Leu), gnomAD 1-155910490-G-T, REVEL 0.67, CADD 23.30
- I42M (p.Ile42Met), rs948974325, Ensembl rs948974325, AlphaMissense 0.78, MetaLR 0.34, Variant assessed as somatic; moderate impact.
- I42T (p.Ile42Thr), rs765636979, ClinGen CA1151881, ClinVar RCV003742312, ClinVar RCV004371872, REVEL 0.68, CADD 25.70, Uncertain significance, Cardiovascular phenotype; Noonan syndrome 8
- S43N (p.Ser43Asn), cosmic curated COSV10085, SIFT 0.07
- S43R (p.Ser43Arg), ExAC rs769063568, gnomAD rs769063568, REVEL 0.50, CADD 24.50
- S43T (p.Ser43Thr), rs1400808611, ClinGen CA342776030, ClinVar RCV003740900, TOPMed rs1400808611, REVEL 0.23, CADD 23.90, Uncertain significance, Noonan syndrome 8
- S43C (p.Ser43Cys), gnomAD 1-155910486-T-A, REVEL 0.69, CADD 25.40
- H44L (p.His44Leu), rs2527197303, ClinGen CA342776020, ClinVar RCV001261140, ClinVar RCV006466157, Uncertain significance, Noonan syndrome 8
- R45G (p.Arg45Gly), rs1316625491, ClinGen CA342776012, ClinVar RCV002585376, ClinVar RCV005622202, REVEL 0.40, CADD 23.90, Uncertain significance, not provided; Noonan syndrome 8
- R45L (p.Arg45Leu), rs1673569021, ClinGen CA342776008, ClinVar RCV001322286, Ensembl rs1673569021, AlphaMissense 0.67, MetaLR 0.27, Uncertain significance, Noonan syndrome 8
- R45Q (p.Arg45Gln), NCI-TCGA Cosmic COSV6416, cosmic curated COSV64166, REVEL 0.14, CADD 23.10, Uncertain significance, Noonan syndrome 8
- P47L (p.Pro47Leu), rs747376042, ClinGen CA1151879, cosmic curated COSV10085, ClinVar RCV001044625, REVEL 0.42, CADD 23.50, Uncertain significance, not specified; Noonan syndrome 8; Cardiovascular phenotype
- P47Q (p.Pro47Gln), cosmic curated COSV10592
- P47S (p.Pro47Ser), Ensembl rs1673568941, SIFT 0.35
- P47T (p.Pro47Thr), rs1673568941, ClinGen CA342775999, ClinVar RCV003581471, REVEL 0.45, CADD 24.50, Uncertain significance, Noonan syndrome 8
- P47P (p.Pro47Pro), rs1057524417, gnomAD 1-155910472-T-C, CADD 10.10
- E48K (p.Glu48Lys), TOPMed rs1165493340, gnomAD rs1165493340, REVEL 0.53, CADD 31.00, Uncertain significance, Noonan syndrome 8
- E48Q (p.Glu48Gln), TOPMed rs1165493340, gnomAD rs1165493340, REVEL 0.47, CADD 27.50
- D49H (p.Asp49His), rs2102590904, ClinGen CA342775985, ClinVar RCV001813692, ClinVar RCV001885298, AlphaMissense 0.86, MetaLR 0.28, Uncertain significance, Noonan syndrome 8; Noonan syndrome and Noonan-related syndrome
- D49V (p.Asp49Val), rs2527197273, ClinGen CA342775981, ClinVar RCV002710425, Uncertain significance, Noonan syndrome 8
- D49E (p.Asp49Glu), gnomAD 1-155910466-A-T, REVEL 0.40, CADD 0.09
- D49N (p.Asp49Asn), gnomAD 1-155910468-C-T, REVEL 0.34, CADD 26.60
- H50D (p.His50Asp), cosmic curated COSV64166, ExAC rs780585553
- H50R (p.His50Arg), Ensembl rs113618684, SIFT 0.02
- H50P (p.His50Pro), gnomAD 1-155910464-T-G, REVEL 0.73, CADD 28.10
- H50N (p.His50Asn), gnomAD 1-155910465-G-T, REVEL 0.71, CADD 29.40
- D51E (p.Asp51Glu), rs1571999275, cosmic curated COSV10611, NCI-TCGA TCGA novel, ClinGen CA342775966, AlphaMissense 0.99, MetaLR 0.28, Uncertain significance, Noonan syndrome 8; not specified
- D51N (p.Asp51Asn), rs869025190, ClinGen CA342775971, ClinVar RCV004517222, REVEL 0.46, AlphaMissense 0.97, Uncertain significance, Cardiovascular phenotype
- D51V (p.Asp51Val), rs2527197242, cosmic curated COSV64167, ClinGen CA342775968, ClinVar RCV001261141, Uncertain significance, Noonan syndrome
- D51Y (p.Asp51Tyr), rs869025190, ClinGen CA353874, cosmic curated COSV10085, ClinVar RCV000207344, AlphaMissense 0.97, MetaLR 0.53, Uncertain significance, Noonan syndrome 8
- P52H (p.Pro52His), cosmic curated COSV10085
- P52L (p.Pro52Leu), rs1673568262, ClinGen CA342775960, cosmic curated COSV64167, ClinVar RCV004517223, REVEL 0.89, CADD 29.20, Uncertain significance, Cardiovascular phenotype
- P52S (p.Pro52Ser), cosmic curated COSV10821, SIFT 0.01
- P52P (p.Pro52Pro), rs1571999270, gnomAD 1-155910457-G-A, CADD 13.60
- P52A (p.Pro52Ala), gnomAD 1-155910459-G-C, REVEL 0.82, CADD 26.20
- I54I (p.Ile54Ile), rs1474550449, gnomAD 1-155910451-A-T, CADD 9.47
- D56Y (p.Asp56Tyr), cosmic curated COSV64171
- D56V (p.Asp56Val), gnomAD 1-155904801-T-A, REVEL 0.86, MetaLR 0.56
- A57G (p.Ala57Gly), rs672601334, ClinGen CA144537, cosmic curated COSV64170, ClinVar RCV000054404, AlphaMissense 0.79, MetaLR 0.52, Pathogenic/Likely pathogenic, Noonan syndrome and Noonan-related syndrome; Cardiovascular phenotype; RIT1-rela
- A57D (p.Ala57Asp), gnomAD 1-155904798-G-T, REVEL 0.74, MetaLR 0.39
- Y58* (p.Tyr58Ter), cosmic curated COSV64171
- Y58C (p.Tyr58Cys), rs2527182416, ClinGen CA342803547, ClinVar RCV002399300, REVEL 0.93, MetaLR 0.73, Uncertain significance, Cardiovascular phenotype
- Y58D (p.Tyr58Asp), rs2527182426, ClinVar RCV004588966, Uncertain significance, not provided
- Y58Y (p.Tyr58Tyr), gnomAD 1-155904794-A-G, CADD 10.60
- Y58H (p.Tyr58His), gnomAD 1-155904796-A-G, REVEL 0.91, MetaLR 0.59
- Y58N (p.Tyr58Asn), gnomAD 1-155904796-A-T, REVEL 0.89, MetaLR 0.67
- K59N (p.Lys59Asn), TOPMed rs1673400156, gnomAD rs1673400156, REVEL 0.44, MetaLR 0.24
- I60I (p.Ile60Ile), gnomAD 1-155904788-G-T, CADD 11.60
- I60T (p.Ile60Thr), gnomAD 1-155904789-A-G, REVEL 0.19, MetaLR 0.06
- I62I (p.Ile62Ile), gnomAD 1-155904782-G-T, CADD 9.75
- I62M (p.Ile62Met), gnomAD 1-155904782-G-C, REVEL 0.48, MetaLR 0.30
- R63C (p.Arg63Cys), cosmic curated COSV64171
- R63H (p.Arg63His), gnomAD rs1673400003, REVEL 0.50, MetaLR 0.38
- I64I (p.Ile64Ile), gnomAD 1-155904776-A-G, CADD 10.90
- I64T (p.Ile64Thr), gnomAD 1-155904777-A-G, REVEL 0.88, MetaLR 0.56
- D66N (p.Asp66Asn), cosmic curated COSV64171, MetaLR 0.18, MetaSVM -0.92
- D66E (p.Asp66Glu), gnomAD 1-155904770-A-T, REVEL 0.26, MetaLR 0.18
- E67* (p.Glu67Ter), NCI-TCGA Cosmic COSV6417, Variant assessed as somatic; high impact.
- E67D (p.Glu67Asp), TOPMed rs1254003235, MetaLR 0.34, MetaSVM -0.45, Likely benign
- E67K (p.Glu67Lys), cosmic curated COSV64171, TOPMed rs746233241, REVEL 0.48, MetaLR 0.27
- E67E (p.Glu67Glu), rs1254003235, gnomAD 1-155904767-C-T, CADD 7.92
- P68P (p.Pro68Pro), gnomAD 1-155904764-A-G, CADD 12.70
- A69D (p.Ala69Asp), rs2527182321, ClinGen CA342803295, ClinVar RCV003741682, Uncertain significance, Noonan syndrome 8
- A69T (p.Ala69Thr), gnomAD rs1673399713, REVEL 0.53, MetaLR 0.40
- N70S (p.Asn70Ser), TOPMed rs1673399593, REVEL 0.38, MetaLR 0.11, Uncertain significance, Cardiovascular phenotype
- N70Y (p.Asn70Tyr), rs1394425355, ClinGen CA342803278, ClinVar RCV001765957, ClinVar RCV001868650, REVEL 0.39, MetaLR 0.22, Uncertain significance, Cardiovascular phenotype; not provided; Noonan syndrome 8
- L71V (p.Leu71Val), rs777167776, ClinGen CA1151861, NCI-TCGA Cosmic COSV6417, cosmic curated COSV64171, REVEL 0.79, MetaLR 0.60, Uncertain significance, Noonan syndrome 8; not provided; Cardiovascular phenotype
- D72N (p.Asp72Asn), cosmic curated COSV10821, MetaLR 0.14, MetaSVM -0.90
- I73N (p.Ile73Asn), cosmic curated COSV10468
- I73S (p.Ile73Ser), cosmic curated COSV64171, MetaLR 0.80, MetaSVM 0.91
- I73V (p.Ile73Val), gnomAD 1-155904751-T-C, REVEL 0.44, MetaLR 0.31
- L74M (p.Leu74Met), cosmic curated COSV64172, Uncertain significance, not provided
- L74L (p.Leu74Leu), rs1477866832, gnomAD 1-155904746-C-T, CADD 14.30
- D75G (p.Asp75Gly), gnomAD 1-155904744-T-C, REVEL 0.95, MetaLR 0.93
- T76S (p.Thr76Ser), cosmic curated COSV10085, MetaLR 0.89, MetaSVM 1.06
- T76K (p.Thr76Lys), gnomAD 1-155904741-G-T, REVEL 0.92, MetaLR 0.89
Public RIT1 analysis runs
- RIT1 analysis run — RIT1 (534 variants) — completed 2026-08-19