PCSK9 (Proprotein convertase subtilisin/kexin type 9) variants and mutations
PCSK9 (also known as Proprotein convertase subtilisin/kexin type 9) is a human protein-coding gene encoding a proprotein convertase subtilisin/kexin type 9 protein. By binding hepatic LDL receptors and promoting their lysosomal degradation, it reduces receptor recycling and raises circulating LDL cholesterol. Gain-of-function variants cause autosomal dominant hypercholesterolemia, whereas loss-of-function variants lower LDL cholesterol and cardiovascular risk. This analysis covers 1,359 PCSK9 variants and mutations. Of these, 98% have computational variant effect predictions. Disease context includes familial hypercholesterolemia, Hypercholesterolemia, and hypercholesterolemia, autosomal dominant, 3. Example PCSK9 variants include M1R, G2D, and G2S.
Variant analysis overview
- Gene: PCSK9
- Protein: Proprotein convertase subtilisin/kexin type 9
- UniProt accession: Q8NBP7
- Organism: Homo sapiens
- Variants analyzed: 1359
- Variant scope: all variants
- Completed: 2026-05-15
Variant and mutation evidence
- Variant composition: 1,074 unspecified-consequence records; 130 missense variants; 106 synonymous variants; 8 in-frame deletions; 4 in-frame insertions; 20 frameshift variants; 10 stop-gained variants; 2 splice-region variants; 5 substitution
- Prediction scores: 1,336 variants have prediction scores (98% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: familial hypercholesterolemia, Hypercholesterolemia, hypercholesterolemia, autosomal dominant, 3, cardiovascular disease, coronary artery disease, metabolic disease, homozygous familial hypercholesterolemia, Disorder of lipid metabolism, hyperlipidemia, myocardial infarction, atherosclerosis, hypercholesterolemia, familial, 1.
Protein structure and variant hotspots
- Protein features: 2 domains; 4 post-translational modification sites.
- Structural context: 652 variants have structural context.
- PTM context: 9 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, PharmGKB, MaveDB, LitVar.
Notable PCSK9 variants
Examples include M1R, G2D, G2S, G2C, G2V, G2G, T3I, T3N. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1R (p.Met1Arg), rs1209186979, ClinGen CA340482584, ClinVar RCV001178472, ClinVar RCV004807333, ESM-1b 1.00, AlphaMissense 0.12, Uncertain significance, Familial hypercholesterolemia; Hypercholesterolemia, autosomal dominant, 3
- G2D (p.Gly2Asp), rs1018576699, ClinGen CA22791777, ClinVar RCV004007994, gnomAD rs1018576699, REVEL 0.17, ESM-1b 0.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- G2S (p.Gly2Ser), rs2523162641, ClinGen CA340482588, ClinVar RCV004014563, REVEL 0.09, ESM-1b 0.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- G2C (p.Gly2Cys), gnomAD 1-55039841-G-T, REVEL 0.25, ESM-1b 0.62
- G2V (p.Gly2Val), gnomAD 1-55039842-G-T, REVEL 0.28, ESM-1b 0.00
- G2G (p.Gly2Gly), gnomAD 1-55039843-C-A, CADD 7.43
- T3I (p.Thr3Ile), rs966100677, ClinGen CA340482597, ClinVar RCV004012902, ClinVar RCV005403372, REVEL 0.06, ESM-1b 0.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3; Familial hypercholesterolemia
- T3N (p.Thr3Asn), rs966100677, ClinGen CA22791778, ClinVar RCV001968859, TOPMed rs966100677, ESM-1b 0.41, AlphaMissense 0.09, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- T3T (p.Thr3Thr), rs1465865735, gnomAD 1-55039846-C-T, CADD 6.99
- V4F (p.Val4Phe), 1000Genomes rs186669805, ExAC rs186669805, TOPMed rs186669805, gnomAD rs186669805, REVEL 0.03, ESM-1b 0.00, Likely benign
- V4I (p.Val4Ile), rs186669805, ClinGen CA035116, ClinVar RCV000583160, ClinVar RCV000771578, REVEL 0.35, ESM-1b 0.00, Conflicting interpretations, Familial hypercholesterolemia; not specified; Cardiovascular phenotype
- V4L (p.Val4Leu), rs186669805, ClinGen CA340482598, ClinVar RCV001179974, 1000Genomes rs186669805, ESM-1b 0.00, AlphaMissense 0.10, Uncertain significance, Familial hypercholesterolemia
- V4V (p.Val4Val), gnomAD 1-55039849-C-T, CADD 8.42
- S5T (p.Ser5Thr), gnomAD 1-55039851-G-C, REVEL 0.06, ESM-1b 0.00
- S5N (p.Ser5Asn), gnomAD 1-55039851-G-A, REVEL 0.09, ESM-1b 0.76
- S5S (p.Ser5Ser), gnomAD 1-55039852-C-T, CADD 8.56
- S6F (p.Ser6Phe), rs1644584130, ClinGen CA340482615, ClinVar RCV001188804, Ensembl rs1644584130, ESM-1b 0.00, AlphaMissense 0.10, Uncertain significance, Familial hypercholesterolemia
- S6T (p.Ser6Thr), gnomAD 1-55039853-T-A, REVEL 0.04, ESM-1b 0.00
- S6Y (p.Ser6Tyr), gnomAD 1-55039854-C-A, REVEL 0.17, ESM-1b 1.00
- S6S (p.Ser6Ser), gnomAD 1-55039855-C-A, CADD 7.96
- R7G (p.Arg7Gly), ExAC rs772165799, gnomAD rs772165799, REVEL 0.07, ESM-1b 0.00
- R7R (p.Arg7Arg), gnomAD 1-55039856-A-C, CADD 6.34
- R8L (p.Arg8Leu), Ensembl rs1021280547, REVEL 0.07, ESM-1b 0.00, Uncertain significance
- R8Q (p.Arg8Gln), rs1021280547, ClinGen CA22791797, ClinVar RCV003606870, Ensembl rs1021280547, REVEL 0.02, ESM-1b 0.31, Conflicting interpretations, Familial hypercholesterolemia; Hypercholesterolemia, autosomal dominant, 3
- R8W (p.Arg8Trp), rs1426361407, ClinGen CA340482623, ClinVar RCV000772311, ClinVar RCV003605680, REVEL 0.05, ESM-1b 0.00, Uncertain significance, Familial hypercholesterolemia; Hypercholesterolemia, autosomal dominant, 3
- R8R (p.Arg8Arg), gnomAD 1-55039859-C-A, CADD 7.08
- R8P (p.Arg8Pro), gnomAD 1-55039860-G-C, REVEL 0.09, ESM-1b 0.00
- S9F (p.Ser9Phe), gnomAD rs1168829435, ESM-1b 0.00, AlphaMissense 0.09
- S9Y (p.Ser9Tyr), gnomAD 1-55039863-C-A, REVEL 0.09, ESM-1b 0.88
- S9S (p.Ser9Ser), rs562480265, gnomAD 1-55039864-C-T, CADD 7.24
- W10* (p.Trp10Ter), NCI-TCGA TCGA novel, CADD 35.00, Variant assessed as somatic; high impact.
- W10R (p.Trp10Arg), gnomAD 1-55039865-T-A, REVEL 0.11, ESM-1b 0.00
- W10S (p.Trp10Ser), gnomAD 1-55039866-G-C, REVEL 0.05, ESM-1b 0.00
- W11* (p.Trp11Ter), gnomAD rs1164872643, CADD 36.00
- W11L (p.Trp11Leu), gnomAD 1-55039869-G-T, REVEL 0.16, ESM-1b 0.00
- P12L (p.Pro12Leu), rs760558712, ClinGen CA041578, ClinVar RCV001190679, ClinVar RCV001225860, REVEL 0.03, ESM-1b 0.00, Conflicting interpretations, not specified; Hypercholesterolemia, autosomal dominant, 3; Cardiovascular pheno
- P12T (p.Pro12Thr), rs968023760, ClinGen CA22791800, ClinVar RCV001182227, ClinVar RCV002451377, REVEL 0.07, ESM-1b 0.00, Uncertain significance, Cardiovascular phenotype; not specified; Familial hypercholesterolemia
- P12S (p.Pro12Ser), gnomAD 1-55039871-C-T, REVEL 0.07, ESM-1b 0.00
- P12Q (p.Pro12Gln), gnomAD 1-55039872-C-A, REVEL 0.06, ESM-1b 0.00
- P12P (p.Pro12Pro), rs1202453511, gnomAD 1-55039873-G-A, CADD 3.25
- L13M (p.Leu13Met), gnomAD 1-55039874-C-A, REVEL 0.17, ESM-1b 1.00
- L13L (p.Leu13Leu), gnomAD 1-55039876-G-A, CADD 7.47
- P14L (p.Pro14Leu), Ensembl rs201184195, REVEL 0.08, ESM-1b 0.00
- P14S (p.Pro14Ser), rs1644584325, ClinGen CA340482660, ClinVar RCV001182804, ClinVar RCV004008326, REVEL 0.04, ESM-1b 0.00, Uncertain significance, Familial hypercholesterolemia; Hypercholesterolemia, autosomal dominant, 3
- P14P (p.Pro14Pro), gnomAD 1-55039879-A-C, CADD 4.76
- p.Pro14 Leu15insMetLeu, rs371488778, gnomAD 1-55039879-A-AATG, CADD 7.81
- L15M (p.Leu15Met), gnomAD 1-55039880-C-A, REVEL 0.18, ESM-1b 1.00
- L15L (p.Leu15Leu), gnomAD 1-55039882-G-T, CADD 5.35
- L16P (p.Leu16Pro), NCI-TCGA Cosmic COSV5616, REVEL 0.17, ESM-1b 0.00, Variant assessed as somatic; moderate impact.
- L16L (p.Leu16Leu), gnomAD 1-55039883-C-T, CADD 6.48
- p.Leu17 Leu18insMet, rs2100250994, gnomAD 1-55039886-C-CTGA, CADD 14.60
- L18M (p.Leu18Met), ESP rs373295327, TOPMed rs373295327, gnomAD rs373295327, REVEL 0.28, ESM-1b 1.00, Likely benign
- L18R (p.Leu18Arg), rs1322134519, ClinGen CA340482682, ClinVar RCV004016999, TOPMed rs1322134519, REVEL 0.43, ESM-1b 1.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- L18L (p.Leu18Leu), rs373295327, gnomAD 1-55039889-C-T, CADD 8.24
- L19L (p.Leu19Leu), gnomAD 1-55039892-C-T, CADD 7.90
- L19R (p.Leu19Arg), gnomAD 1-55039893-T-G, REVEL 0.46, ESM-1b 1.00
- L20L (p.Leu20Leu), rs1644584779, gnomAD 1-55039897-G-A, CADD 6.36
- p.Leu21 Leu23del, rs1644584450, gnomAD 1-55039878-CACTGC, CADD 14.20
- L21L (p.Leu21Leu), rs1644584793, gnomAD 1-55039898-C-T, CADD 7.74
- L22F (p.Leu22Phe), TOPMed rs1266907594, gnomAD rs1266907594, REVEL 0.19, ESM-1b 1.00
- L22P (p.Leu22Pro), rs1644584917, ClinGen CA340482704, ClinVar RCV001190098, ClinVar RCV004010409, REVEL 0.38, ESM-1b 0.13, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3; Cardiovascular phenotype; Familial
- p.Leu22 Leu23del, rs35574083, gnomAD 1-55039879-ACTGCT, CADD 9.59
- L22I (p.Leu22Ile), gnomAD 1-55039901-C-A, REVEL 0.11, ESM-1b 1.00
- L22L (p.Leu22Leu), gnomAD 1-55039903-C-A, CADD 7.66
- L23R (p.Leu23Arg), TOPMed rs1557497443, REVEL 0.35, ESM-1b 0.00
- L23del (p.Leu23del), rs1453893690, gnomAD 1-55039878-CACT-C, CADD 7.46
- p.Leu23dup, rs35574083, gnomAD 1-55039879-A-ACTG, CADD 7.93
- L23P (p.Leu23Pro), gnomAD 1-55039902-T-TG, CADD 23.50
- L23S (p.Leu23Ser), gnomAD 1-55039903-C-CT, CADD 22.00
- L23F (p.Leu23Phe), gnomAD 1-55039903-C-CTT, CADD 21.70
- L23L (p.Leu23Leu), gnomAD 1-55039906-G-T, CADD 8.85
- G24A (p.Gly24Ala), gnomAD rs1183261419, REVEL 0.04, ESM-1b 0.00
- G24C (p.Gly24Cys), rs1479030404, ClinGen CA340482713, ClinVar RCV004014634, REVEL 0.06, ESM-1b 0.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- G24S (p.Gly24Ser), rs1479030404, ClinGen CA340482711, ClinVar RCV001190241, ClinVar RCV003163473, REVEL 0.06, ESM-1b 0.00, Uncertain significance, Cardiovascular phenotype; Familial hypercholesterolemia; Hypercholesterolemia, a
- G24D (p.Gly24Asp), gnomAD 1-55039908-G-A, REVEL 0.06, ESM-1b 0.80
- G24G (p.Gly24Gly), gnomAD 1-55039909-T-G, CADD 3.17
- P25A (p.Pro25Ala), ExAC rs776276715, TOPMed rs776276715, gnomAD rs776276715, REVEL 0.19, ESM-1b 0.00, Likely benign, Familial hypercholesterolemia
- P25L (p.Pro25Leu), TOPMed rs1247850588, gnomAD rs1247850588, REVEL 0.19, ESM-1b 0.00
- P25S (p.Pro25Ser), ExAC rs776276715, TOPMed rs776276715, gnomAD rs776276715, REVEL 0.23, ESM-1b 0.00
- P25T (p.Pro25Thr), gnomAD 1-55039910-C-A, REVEL 0.25, ESM-1b 0.00
- P25P (p.Pro25Pro), gnomAD 1-55039912-C-A, CADD 5.74
- A26R (p.Ala26Arg), rs775052433, ClinGen CA044217, ClinVar RCV004016923, Likely benign
- A26T (p.Ala26Thr), rs1553135400, ClinGen CA340482722, ClinVar RCV000508903, ClinVar RCV004023448, REVEL 0.03, ESM-1b 0.00, Uncertain significance, Cardiovascular phenotype; not specified
- A26V (p.Ala26Val), rs1413443246, ClinGen CA340482727, ClinVar RCV001183762, ClinVar RCV002411693, REVEL 0.06, ESM-1b 0.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3; Cardiovascular phenotype
- A26S (p.Ala26Ser), gnomAD 1-55039913-G-T, REVEL 0.03, ESM-1b 0.00
- A26P (p.Ala26Pro), gnomAD 1-55039913-G-C, REVEL 0.06, ESM-1b 0.00
- A26E (p.Ala26Glu), gnomAD 1-55039914-C-A, REVEL 0.04, ESM-1b 0.00
- A26A (p.Ala26Ala), gnomAD 1-55039915-G-T, CADD 1.52
- G27A (p.Gly27Ala), rs1187613601, ClinGen CA340482732, ClinVar RCV001178695, TOPMed rs1187613601, ESM-1b 0.00, AlphaMissense 0.07, Uncertain significance, Familial hypercholesterolemia
- G27D (p.Gly27Asp), rs1187613601, ClinGen CA340482731, ClinVar RCV002419483, ClinVar RCV003581847, REVEL 0.11, ESM-1b 1.00, Uncertain significance, Cardiovascular phenotype; Familial hypercholesterolemia; not specified
- G27S (p.Gly27Ser), TOPMed rs1644585224, gnomAD rs1644585224, REVEL 0.04, ESM-1b 0.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- G27V (p.Gly27Val), TOPMed rs1187613601, gnomAD rs1187613601, REVEL 0.04, ESM-1b 0.00, Uncertain significance, Cardiovascular phenotype
- G27R (p.Gly27Arg), gnomAD 1-55039914-CGG-C, CADD 16.80
- G27C (p.Gly27Cys), gnomAD 1-55039916-G-T, REVEL 0.13, ESM-1b 0.22
- G27G (p.Gly27Gly), gnomAD 1-55039918-C-A, CADD 5.23
- A28S (p.Ala28Ser), NCI-TCGA TCGA novel, REVEL 0.05, ESM-1b 0.00, Variant assessed as somatic; moderate impact.
- A28T (p.Ala28Thr), rs547860327, ClinGen CA044814, ClinVar RCV004016349, 1000Genomes rs547860327, REVEL 0.05, ESM-1b 0.00, Uncertain significance, not specified; Hypercholesterolemia, autosomal dominant, 3; Cardiovascular pheno
- A28D (p.Ala28Asp), gnomAD 1-55039920-C-A, REVEL 0.09, ESM-1b 0.77
- R29C (p.Arg29Cys), rs866597555, ClinGen CA340482740, ClinVar RCV001179816, gnomAD rs866597555, REVEL 0.11, ESM-1b 0.62, Uncertain significance, Familial hypercholesterolemia
- R29G (p.Arg29Gly), rs866597555, ClinGen CA340482739, ClinVar RCV001097310, ClinVar RCV001097311, ESM-1b 0.00, AlphaMissense 0.16, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3; Hypobetalipoproteinemia
- R29H (p.Arg29His), rs1160058809, ClinGen CA340482741, ClinVar RCV002998883, ClinVar RCV004065232, REVEL 0.11, ESM-1b 0.51, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3; Cardiovascular phenotype; not provi
- R29P (p.Arg29Pro), TOPMed rs1160058809, gnomAD rs1160058809, REVEL 0.05, ESM-1b 0.00, Uncertain significance
- R29S (p.Arg29Ser), gnomAD rs866597555, REVEL 0.03, ESM-1b 0.00, Uncertain significance
- R29V (p.Arg29Val), rs1553135406, gnomAD 1-55039919-GC-G, CADD 18.40
- R29L (p.Arg29Leu), gnomAD 1-55039923-G-T, REVEL 0.03, ESM-1b 0.00
- A30E (p.Ala30Glu), rs958750957, ClinGen CA340482747, ClinVar RCV001187942, gnomAD rs958750957, REVEL 0.23, ESM-1b 0.40, Uncertain significance, Familial hypercholesterolemia
- A30G (p.Ala30Gly), gnomAD rs958750957, REVEL 0.20, ESM-1b 0.00, Uncertain significance
- A30T (p.Ala30Thr), gnomAD 1-55039925-G-A, REVEL 0.14, ESM-1b 0.00
- A30S (p.Ala30Ser), gnomAD 1-55039925-G-T, REVEL 0.08, ESM-1b 0.00
- A30V (p.Ala30Val), gnomAD 1-55039926-C-T, REVEL 0.21, ESM-1b 0.00
- A30A (p.Ala30Ala), rs1644585418, gnomAD 1-55039927-G-A, CADD 8.73
- Q31E (p.Gln31Glu), gnomAD rs1304809659, REVEL 0.05, ESM-1b 0.00, Uncertain significance, Familial hypercholesterolemia
- Q31H (p.Gln31His), rs1344705474, gnomAD 1-55039925-G-GCGC, CADD 22.80
- Q31K (p.Gln31Lys), gnomAD 1-55039928-C-A, REVEL 0.06, ESM-1b 0.10
- Q31* (p.Gln31Ter), gnomAD 1-55039928-C-T, CADD 35.00
- Q31R (p.Gln31Arg), gnomAD 1-55039929-A-G, REVEL 0.17, ESM-1b 0.00
- E32D (p.Glu32Asp), rs1291205662, ClinGen CA340482762, ClinVar RCV004012885, ESM-1b 0.00, AlphaMissense 0.10, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- E32K (p.Glu32Lys), rs564427867, ClinGen CA045184, ClinVar RCV000331053, ClinVar RCV000775016, REVEL 0.43, ESM-1b 0.47, Pathogenic/Likely pathogenic, Homozygous familial hypercholesterolemia; Hypercholesterolemia, autosomal domina
- E32Q (p.Glu32Gln), gnomAD 1-55039931-G-C, REVEL 0.07, ESM-1b 0.00
- E32G (p.Glu32Gly), gnomAD 1-55039932-A-G, REVEL 0.05, ESM-1b 0.00
- E32E (p.Glu32Glu), rs1291205662, gnomAD 1-55039933-G-A, CADD 4.26
- D33N (p.Asp33Asn), rs917219621, ClinGen CA22792017, ClinVar RCV001190553, ClinVar RCV001876229, REVEL 0.17, ESM-1b 0.86, Uncertain significance, Familial hypercholesterolemia; Hypercholesterolemia, autosomal dominant, 3; not
- D33E (p.Asp33Glu), gnomAD 1-55039936-C-G, REVEL 0.06, ESM-1b 0.00
- D33D (p.Asp33Asp), gnomAD 1-55039936-C-T, CADD 7.63
- E34K (p.Glu34Lys), rs371030381, ClinGen CA034587, ClinVar RCV000644532, ClinVar RCV000775253, REVEL 0.04, ESM-1b 0.68, Uncertain significance, Hypobetalipoproteinemia; Cardiovascular phenotype; not specified
- E34* (p.Glu34Ter), gnomAD 1-55039937-G-T, CADD 37.00
- E34G (p.Glu34Gly), gnomAD 1-55039938-A-G, REVEL 0.04, ESM-1b 0.00
- E34D (p.Glu34Asp), gnomAD 1-55039939-G-T, REVEL 0.07, ESM-1b 0.00
- D35G (p.Asp35Gly), NCI-TCGA TCGA novel, REVEL 0.19, ESM-1b 0.00, Variant assessed as somatic; moderate impact.
- D35Y (p.Asp35Tyr), rs764603059, ClinGen CA034785, ClinVar RCV000417231, ClinVar RCV000775254, REVEL 0.32, ESM-1b 0.00, Conflicting interpretations, PCSK9-related disorder; Cardiovascular phenotype; Familial hypercholesterolemia
- D35R (p.Asp35Arg), gnomAD 1-55039938-AGGACG, CADD 23.80
- D35H (p.Asp35His), gnomAD 1-55039940-G-C, REVEL 0.19, ESM-1b 0.54
- D35D (p.Asp35Asp), rs533474523, gnomAD 1-55039942-C-T, CADD 7.82
- G36C (p.Gly36Cys), ExAC rs757753730, TOPMed rs757753730, gnomAD rs757753730, REVEL 0.15, ESM-1b 0.84, Uncertain significance
- G36D (p.Gly36Asp), rs1256244941, ClinGen CA340482787, ClinVar RCV003172697, ClinVar RCV004808459, REVEL 0.05, ESM-1b 0.00, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3; Cardiovascular phenotype
- G36S (p.Gly36Ser), rs757753730, ClinGen CA034887, ClinVar RCV001181022, ClinVar RCV001321345, REVEL 0.05, ESM-1b 0.00, Uncertain significance, Cardiovascular phenotype; Familial hypercholesterolemia; Hypercholesterolemia, a
- G36V (p.Gly36Val), NCI-TCGA TCGA novel, REVEL 0.05, ESM-1b 0.00, Variant assessed as somatic; moderate impact.
- G36R (p.Gly36Arg), gnomAD 1-55039943-G-C, REVEL 0.10, ESM-1b 0.00
- G36G (p.Gly36Gly), gnomAD 1-55039945-C-A, CADD 8.23
- D37E (p.Asp37Glu), rs1210705445, ClinGen CA340482796, ClinVar RCV002437815, ClinVar RCV003481312, REVEL 0.07, ESM-1b 0.00, Uncertain significance, not provided; Hypercholesterolemia, autosomal dominant, 3; Cardiovascular phenot
- D37Y (p.Asp37Tyr), TOPMed rs1360174848, REVEL 0.26, ESM-1b 0.00, Uncertain significance, Familial hypercholesterolemia
- D37N (p.Asp37Asn), gnomAD 1-55039946-G-A, REVEL 0.14, ESM-1b 0.01
- D37G (p.Asp37Gly), gnomAD 1-55039947-A-G, REVEL 0.06, ESM-1b 0.00
- D37D (p.Asp37Asp), rs1210705445, gnomAD 1-55039948-C-T, CADD 10.70
- Y38C (p.Tyr38Cys), rs2523164477, ClinGen CA340482801, ClinVar RCV003500192, REVEL 0.29, ESM-1b 0.66, Uncertain significance, Hypercholesterolemia, autosomal dominant, 3
- Y38H (p.Tyr38His), TOPMed rs971757977, gnomAD rs971757977, REVEL 0.07, ESM-1b 0.00, Uncertain significance, Familial hypercholesterolemia
- Y38F (p.Tyr38Phe), gnomAD 1-55039950-A-T, REVEL 0.04, ESM-1b 0.00
- Y38* (p.Tyr38Ter), gnomAD 1-55039951-C-G, CADD 36.00
- Y38Y (p.Tyr38Tyr), gnomAD 1-55039951-C-T, CADD 10.70
- E39K (p.Glu39Lys), rs781590513, ClinGen CA035375, ClinVar RCV001181023, ClinVar RCV001876014, REVEL 0.15, ESM-1b 0.25, Uncertain significance, Familial hypercholesterolemia; Hypercholesterolemia, autosomal dominant, 3
- E39V (p.Glu39Val), Ensembl rs1644585712, REVEL 0.21, ESM-1b 0.00
- E39* (p.Glu39Ter), gnomAD 1-55039952-G-T, CADD 37.00
- E39Q (p.Glu39Gln), gnomAD 1-55039952-G-C, REVEL 0.12, ESM-1b 0.00
- E39D (p.Glu39Asp), gnomAD 1-55039954-G-T, REVEL 0.03, ESM-1b 0.00
- E39E (p.Glu39Glu), gnomAD 1-55039954-G-A, CADD 12.40
- E40K (p.Glu40Lys), rs1416330878, ClinGen CA340482812, ClinVar RCV001057193, ClinVar RCV003581771, REVEL 0.10, ESM-1b 0.00, Conflicting interpretations, Cardiovascular phenotype; not provided; Hypercholesterolemia, autosomal dominant
- E40* (p.Glu40Ter), gnomAD 1-55039955-G-T, CADD 44.00
- E40G (p.Glu40Gly), gnomAD 1-55039956-A-G, REVEL 0.07, ESM-1b 0.00
- E40D (p.Glu40Asp), gnomAD 1-55039957-G-T, REVEL 0.06, ESM-1b 0.00
- E40E (p.Glu40Glu), gnomAD 1-55039957-G-A, CADD 13.30
- L41Q (p.Leu41Gln), rs550263135, ClinGen CA036030, ClinVar RCV003305370, ClinVar RCV003500823, REVEL 0.41, ESM-1b 0.00, Uncertain significance, Cardiovascular phenotype; not specified; Hypercholesterolemia, autosomal dominan
- L41V (p.Leu41Val), ExAC rs770290145, gnomAD rs770290145, REVEL 0.08, ESM-1b 0.00
- L41L (p.Leu41Leu), gnomAD 1-55039958-C-T, CADD 13.20
- L41M (p.Leu41Met), gnomAD 1-55039958-C-A, REVEL 0.12, ESM-1b 0.00
- L41P (p.Leu41Pro), gnomAD 1-55039959-T-C, REVEL 0.39, ESM-1b 0.00
- V42M (p.Val42Met), gnomAD 1-55039961-G-A, REVEL 0.05, ESM-1b 0.00
- V42V (p.Val42Val), rs374142123, gnomAD 1-55039963-G-T, CADD 11.10
- L43L (p.Leu43Leu), gnomAD 1-55039964-C-T, CADD 10.80
- L43I (p.Leu43Ile), gnomAD 1-55039964-C-A, REVEL 0.23, ESM-1b 0.37
- L43P (p.Leu43Pro), gnomAD 1-55039965-T-C, REVEL 0.47, ESM-1b 0.00
- A44G (p.Ala44Gly), Ensembl rs1644585825, REVEL 0.05, ESM-1b 0.00
- A44S (p.Ala44Ser), Ensembl rs773660398, REVEL 0.06, ESM-1b 0.00
- A44T (p.Ala44Thr), Ensembl rs773660398, REVEL 0.06, ESM-1b 0.00
- A44V (p.Ala44Val), gnomAD 1-55039968-C-T, REVEL 0.04, ESM-1b 0.00
- A44D (p.Ala44Asp), gnomAD 1-55039968-C-A, REVEL 0.28, ESM-1b 0.00
- A44A (p.Ala44Ala), rs1178309760, gnomAD 1-55039969-C-G, CADD 12.50
- L45S (p.Leu45Ser), gnomAD rs1360032511, REVEL 0.34, ESM-1b 0.00
- L45L (p.Leu45Leu), rs2100252140, gnomAD 1-55039970-T-C, CADD 13.50
- L45V (p.Leu45Val), gnomAD 1-55039970-T-G, REVEL 0.11, ESM-1b 0.00
- L45M (p.Leu45Met), gnomAD 1-55039970-T-A, REVEL 0.18, ESM-1b 0.00
Public PCSK9 analysis runs
- PCSK9 analysis run — PCSK9 (1,359 variants) — completed 2026-05-15