CDH2 (Cadherin-2) variants and mutations
CDH2 (also known as Cadherin-2) is a human protein-coding gene encoding a cadherin-2 protein. It mediates calcium-dependent cell-cell adhesion in neural, cardiac, and mesenchymal tissues and helps organize adherens junctions during development. Heterozygous pathogenic variants can cause a syndromic neurodevelopmental disorder with variable cardiac and craniofacial abnormalities. This analysis covers 1,342 CDH2 variants and mutations. Of these, 86% have computational variant effect predictions. Disease context includes agenesis of corpus callosum, cardiac, ocular, and genital syndrome, arrhythmogenic right ventricular dysplasia, familial, 14, and Agenesis of corpus callosum. Example CDH2 variants include R3G, R3Q, and R3W.
Variant analysis overview
- Gene: CDH2
- Protein: Cadherin-2
- UniProt accession: P19022
- Organism: Homo sapiens
- Variants analyzed: 1342
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 1,178 unspecified-consequence records; 1 stop retained variant; 73 synonymous variants; 74 missense variants; 2 stop lost; 3 in-frame deletions; 3 splice-region variants; 4 frameshift variants; 1 stop-gained variants; 1 in-frame insertions; 2 substitution
- Prediction scores: 1,155 variants have prediction scores (86% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: agenesis of corpus callosum, cardiac, ocular, and genital syndrome, arrhythmogenic right ventricular dysplasia, familial, 14, Agenesis of corpus callosum, attention deficit-hyperactivity disorder 8, familial isolated arrhythmogenic ventricular dysplasia, right dominant form, neurodegenerative disease, auditory neuropathy, aortic valve disorder, mathematical ability, ventricular fibrillation, placental retention, Abnormality of refraction.
Protein structure and variant hotspots
- Protein features: 1 transmembrane segments; 5 domains; 15 binding sites; 9 post-translational modification sites.
- Structural context: 772 variants have structural context.
- PTM context: 8 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable CDH2 variants
Examples include R3G, R3Q, R3W, I4R, A5V, A7G, A7T, A7V. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- R3G (p.Arg3Gly), ExAC rs761151029, TOPMed rs761151029, gnomAD rs761151029, REVEL 0.28, MetaLR 0.09
- R3Q (p.Arg3Gln), rs1323181717, ClinGen CA402245147, ClinVar RCV002016860, ClinVar RCV002372805, REVEL 0.21, MetaLR 0.09, Uncertain significance, not provided; Inborn genetic diseases
- R3W (p.Arg3Trp), ExAC rs761151029, TOPMed rs761151029, gnomAD rs761151029, REVEL 0.19, MetaLR 0.09, Uncertain significance, not provided
- I4R (p.Ile4Arg), rs2510801382, ClinGen CA402245141, ClinVar RCV002994842, ClinVar RCV004801267, Uncertain significance, not specified; not provided
- A5V (p.Ala5Val), rs1284853215, ClinGen CA402245134, ClinVar RCV002227796, ClinVar RCV002391374, REVEL 0.06, MetaLR 0.07, Conflicting interpretations, Arrhythmogenic right ventricular dysplasia, familial, 14; not provided; Inborn g
- A7G (p.Ala7Gly), TOPMed rs1598530655, REVEL 0.20, MetaLR 0.12
- A7T (p.Ala7Thr), Ensembl rs1568028773, REVEL 0.21, MetaLR 0.12
- A7V (p.Ala7Val), TOPMed rs1598530655, REVEL 0.24, MetaLR 0.10
- L8P (p.Leu8Pro), rs1293733346, ClinGen CA402245119, ClinVar RCV002430671, ClinVar RCV005058786, REVEL 0.15, MetaLR 0.07, Conflicting interpretations, Inborn genetic diseases; not provided
- L8V (p.Leu8Val), rs1369360558, ClinGen CA402245120, ClinVar RCV002446301, TOPMed rs1369360558, REVEL 0.11, MetaLR 0.08, Uncertain significance, Inborn genetic diseases
- R9G (p.Arg9Gly), rs1403830213, ClinGen CA402245116, ClinVar RCV002745226, 1000Genomes rs1403830213, REVEL 0.29, MetaLR 0.06, Uncertain significance, not provided
- R9Q (p.Arg9Gln), 1000Genomes rs2144382434, REVEL 0.19, MetaLR 0.05
- R9W (p.Arg9Trp), 1000Genomes rs1403830213, TOPMed rs1403830213, gnomAD rs1403830213, REVEL 0.16, MetaLR 0.09, Uncertain significance, not provided
- T10A (p.Thr10Ala), rs879030779, ClinGen CA297936936, ClinVar RCV001889396, ClinVar RCV005535106, REVEL 0.06, MetaLR 0.07, Uncertain significance, Inborn genetic diseases; not provided
- T10I (p.Thr10Ile), rs773400550, ClinGen CA402245108, ClinVar RCV002435606, ClinVar RCV003102961, REVEL 0.12, MetaLR 0.07, Uncertain significance, Inborn genetic diseases; not provided
- T10N (p.Thr10Asn), rs773400550, ClinGen CA8923863, ClinVar RCV002622553, ClinVar RCV005535372, REVEL 0.14, MetaLR 0.07, Uncertain significance, Inborn genetic diseases; not provided
- T10P (p.Thr10Pro), rs879030779, ClinGen CA402245110, ClinVar RCV002438031, ClinVar RCV003102852, REVEL 0.23, MetaLR 0.07, Uncertain significance, Inborn genetic diseases; not provided
- T10S (p.Thr10Ser), rs879030779, ClinGen CA402245111, ClinVar RCV002649760, ClinVar RCV003308200, REVEL 0.14, MetaLR 0.07, Uncertain significance, Inborn genetic diseases; not provided
- L11V (p.Leu11Val), rs1351191506, ClinGen CA402245106, ClinVar RCV002707901, NCI-TCGA TCGA novel, Uncertain significance, Inborn genetic diseases
- L12R (p.Leu12Arg), Ensembl rs2016555703
- P13L (p.Pro13Leu), TOPMed rs1363152842, gnomAD rs1363152842, REVEL 0.28, MetaLR 0.11
- P13S (p.Pro13Ser), rs1420154381, ClinGen CA402245096, ClinVar RCV002028278, ClinVar RCV002361365, REVEL 0.22, MetaLR 0.10, Uncertain significance, not provided; Inborn genetic diseases
- L14P (p.Leu14Pro), rs1434663670, ClinGen CA402245084, ClinVar RCV003704784, gnomAD rs1434663670, REVEL 0.30, MetaLR 0.15, Uncertain significance, not provided
- A16T (p.Ala16Thr), rs1456038030, ClinGen CA402245070, ClinVar RCV002743710, Ensembl rs1456038030, REVEL 0.16, MetaLR 0.10, Uncertain significance, Inborn genetic diseases
- A16V (p.Ala16Val), TOPMed rs1490213867, gnomAD rs1490213867, REVEL 0.21, MetaLR 0.09
- A17V (p.Ala17Val), rs1219438806, ClinGen CA402245052, ClinVar RCV003857978, TOPMed rs1219438806, REVEL 0.22, MetaLR 0.09, Uncertain significance, not provided
- L19F (p.Leu19Phe), gnomAD rs1214159271, REVEL 0.05, MetaLR 0.08, Uncertain significance, not provided
- L19P (p.Leu19Pro), rs2016554850, ClinGen CA402245036, ClinVar RCV003368152, gnomAD rs2016554850, REVEL 0.26, MetaLR 0.09, Uncertain significance, Inborn genetic diseases
- Q20E (p.Gln20Glu), rs2510801262, ClinGen CA402245031, ClinVar RCV002996894, REVEL 0.19, MetaLR 0.08, Uncertain significance, not provided
- Q20H (p.Gln20His), TOPMed rs1332308156, gnomAD rs1332308156, REVEL 0.22, MetaLR 0.09
- Q20R (p.Gln20Arg), Ensembl rs2144382248, REVEL 0.27, MetaLR 0.08
- A21E (p.Ala21Glu), ExAC rs751608409, TOPMed rs751608409, gnomAD rs751608409, REVEL 0.17, MetaLR 0.09, Uncertain significance
- A21S (p.Ala21Ser), rs17495042, ClinGen CA402244776, ClinVar RCV001876425, 1000Genomes rs17495042, REVEL 0.12, MetaLR 0.09, Uncertain significance, not provided
- A21T (p.Ala21Thr), rs17495042, ClinGen CA8923844, ClinVar RCV002084752, ClinVar RCV005628333, REVEL 0.06, MetaLR 0.03, Benign/Likely benign, not provided; not specified
- A21V (p.Ala21Val), rs751608409, ClinGen CA8923843, ClinVar RCV002368778, ClinVar RCV006470916, REVEL 0.07, MetaLR 0.07, Uncertain significance, Inborn genetic diseases; not provided
- S22C (p.Ser22Cys), Ensembl rs2144327457
- S22F (p.Ser22Phe), Ensembl rs2144327457, REVEL 0.21, MetaLR 0.10
- V23A (p.Val23Ala), rs201041020, ClinGen CA297933416, ClinVar RCV002675941, ClinVar RCV005535386, AlphaMissense 0.05, MetaLR 0.07, Uncertain significance, not provided; Inborn genetic diseases
- V23L (p.Val23Leu), ExAC rs755151089, gnomAD rs755151089, REVEL 0.11, MetaLR 0.06
- E24Q (p.Glu24Gln), rs146386375, ClinGen CA8923840, ClinVar RCV001985159, ClinVar RCV003170102, REVEL 0.08, MetaLR 0.07, Conflicting interpretations, Inborn genetic diseases; not provided
- A25S (p.Ala25Ser), rs2510778357, ClinGen CA402244740, ClinVar RCV003231736, Uncertain significance, not provided
- A25T (p.Ala25Thr), rs2510778357, ClinGen CA402244742, ClinVar RCV003709140, REVEL 0.22, MetaLR 0.18, Uncertain significance, not provided
- S26F (p.Ser26Phe), ExAC rs766647206, gnomAD rs766647206, REVEL 0.15, MetaLR 0.08
- G27C (p.Gly27Cys), gnomAD rs1462592216
- G27S (p.Gly27Ser), gnomAD rs1462592216, REVEL 0.13, MetaLR 0.07, Uncertain significance, not provided
- G27V (p.Gly27Val), NCI-TCGA Cosmic COSV5227, MetaLR 0.08, MetaSVM -1.06, Variant assessed as somatic; moderate impact.
- I29N (p.Ile29Asn), rs1372513645, ClinGen CA402244697, ClinVar RCV003021847, ClinVar RCV003358048, REVEL 0.17, MetaLR 0.06, Uncertain significance, Inborn genetic diseases; not provided
- A30T (p.Ala30Thr), rs200711868, ClinGen CA8923837, ClinVar RCV002122537, ExAC rs200711868, REVEL 0.14, MetaLR 0.06, Likely benign, not provided
- C32Y (p.Cys32Tyr), NCI-TCGA TCGA novel, MetaLR 0.67, MetaSVM 0.38, Variant assessed as somatic; moderate impact.
- K33* (p.Lys33Ter), NCI-TCGA Cosmic COSV5228, Variant assessed as somatic; high impact.
- K33E (p.Lys33Glu), rs201462293, ClinGen CA8923835, ClinVar RCV002387226, ClinVar RCV003774212, REVEL 0.12, MetaLR 0.11, Uncertain significance, Inborn genetic diseases; not provided
- K33N (p.Lys33Asn), NCI-TCGA TCGA novel, MetaLR 0.09, MetaSVM -1.06, Uncertain significance, not provided
- P37L (p.Pro37Leu), rs774902934, ClinGen CA8923834, ClinVar RCV002611922, ClinVar RCV003368022, REVEL 0.16, MetaLR 0.06, Uncertain significance, Inborn genetic diseases; not provided
- E38K (p.Glu38Lys), rs1274623800, ClinGen CA402244601, ClinVar RCV002665382, ClinVar RCV003777600, REVEL 0.30, MetaLR 0.21, Uncertain significance, not provided; Inborn genetic diseases
- D39E (p.Asp39Glu), rs879180473, ClinGen CA402244579, ClinVar RCV002653719, TOPMed rs879180473, REVEL 0.24, MetaLR 0.11, Uncertain significance, not provided
- D39G (p.Asp39Gly), ExAC rs769118218, TOPMed rs769118218, gnomAD rs769118218, REVEL 0.21, MetaLR 0.20, Uncertain significance, Inborn genetic diseases
- D39N (p.Asp39Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- D39V (p.Asp39Val), ExAC rs769118218, TOPMed rs769118218, gnomAD rs769118218, REVEL 0.26, MetaLR 0.23, Uncertain significance
- D39Y (p.Asp39Tyr), TOPMed rs2016058289
- V40I (p.Val40Ile), TOPMed rs1197088956
- Y41* (p.Tyr41Ter), ExAC rs757055934, gnomAD rs757055934, CADD 34.00
- V44A (p.Val44Ala), ExAC rs774927665, TOPMed rs774927665, gnomAD rs774927665, REVEL 0.11, MetaLR 0.09
- V44F (p.Val44Phe), gnomAD rs1246347582, REVEL 0.17, MetaLR 0.12
- L45S (p.Leu45Ser), rs2510778265, ClinGen CA402244516, ClinVar RCV002922316, Uncertain significance, not provided
- S46L (p.Ser46Leu), rs780887307, ClinGen CA8923826, ClinVar RCV002676244, ExAC rs780887307, REVEL 0.16, MetaLR 0.09, Uncertain significance, not provided
- S46W (p.Ser46Trp), NCI-TCGA TCGA novel, REVEL 0.24, MetaLR 0.16, Variant assessed as somatic; moderate impact.
- K47R (p.Lys47Arg), rs980711081, []
- D48Y (p.Asp48Tyr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V49M (p.Val49Met), rs2510778241, ClinGen CA402244474, ClinVar RCV003687952, REVEL 0.09, MetaLR 0.13, Uncertain significance, not provided
- H50R (p.His50Arg), rs1026380265, ClinGen CA297933412, ClinVar RCV002389863, ClinVar RCV006470056, REVEL 0.05, MetaLR 0.08, Uncertain significance, not provided; Inborn genetic diseases
- H50Y (p.His50Tyr), rs150672295, ClinGen CA8923823, ClinVar RCV001959661, 1000Genomes rs150672295, REVEL 0.10, MetaLR 0.12, Uncertain significance, not provided
- E51D (p.Glu51Asp), NCI-TCGA Cosmic COSV5227, NCI-TCGA Cosmic COSV9929, MetaLR 0.14, MetaSVM -1.00, Variant assessed as somatic; moderate impact.
- G52* (p.Gly52Ter), NCI-TCGA Cosmic COSV9929, Variant assessed as somatic; high impact.
- G52E (p.Gly52Glu), NCI-TCGA Cosmic COSV5229, Variant assessed as somatic; moderate impact.
- G52R (p.Gly52Arg), NCI-TCGA Cosmic COSV9929, Variant assessed as somatic; moderate impact.
- P54L (p.Pro54Leu), TOPMed rs2016057486, MetaLR 0.11, MetaSVM -1.01
- L56F (p.Leu56Phe), NCI-TCGA Cosmic COSV5228, NCI-TCGA Cosmic COSV5229, REVEL 0.23, MetaLR 0.24, Variant assessed as somatic; moderate impact.
- N57S (p.Asn57Ser), TOPMed rs1459488007, gnomAD rs1459488007, REVEL 0.09, MetaLR 0.10
- K59T (p.Lys59Thr), NCI-TCGA Cosmic COSV5229, cosmic curated COSV52295, REVEL 0.10, MetaLR 0.07, Variant assessed as somatic; moderate impact.
- S61C (p.Ser61Cys), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, Variant assessed as somatic; moderate impact.
- N64H (p.Asn64His), rs202205175, ClinGen CA8923755, ClinVar RCV002016398, 1000Genomes rs202205175, REVEL 0.15, MetaLR 0.12, Uncertain significance, not provided
- N64S (p.Asn64Ser), rs779271742, ClinGen CA8923754, ClinVar RCV002410661, ClinVar RCV005097834, REVEL 0.10, MetaLR 0.07, Uncertain significance, not provided; Inborn genetic diseases
- G65E (p.Gly65Glu), rs1357817564, ClinGen CA402244791, NCI-TCGA Cosmic COSV5228, cosmic curated COSV52280, REVEL 0.11, MetaLR 0.09, Uncertain significance, not provided
- K66E (p.Lys66Glu), ExAC rs201274796, gnomAD rs201274796, REVEL 0.15, MetaLR 0.09, Uncertain significance, not provided
- R67I (p.Arg67Ile), ExAC rs766988186, TOPMed rs766988186, gnomAD rs766988186, REVEL 0.15, MetaLR 0.16, Uncertain significance, Inborn genetic diseases; not provided
- K68I (p.Lys68Ile), rs2013168180, ClinGen CA402244749, ClinVar RCV002646936, TOPMed rs2013168180, AlphaMissense 0.16, MetaLR 0.17, Uncertain significance, not provided
- V69I (p.Val69Ile), cosmic curated COSV52275, ExAC rs755723588, TOPMed rs755723588, gnomAD rs755723588, REVEL 0.07, MetaLR 0.04
- Q70E (p.Gln70Glu), rs1372835307, ClinGen CA402244724, ClinVar RCV002424015, ClinVar RCV005097935, REVEL 0.08, MetaLR 0.10, Uncertain significance, Inborn genetic diseases; not provided
- E72D (p.Glu72Asp), NCI-TCGA Cosmic COSV5227, cosmic curated COSV52278, REVEL 0.17, MetaLR 0.11, Variant assessed as somatic; moderate impact.
- E72K (p.Glu72Lys), rs1290280143, ClinGen CA402244686, ClinVar RCV002726614, TOPMed rs1290280143, REVEL 0.16, MetaLR 0.16, Uncertain significance, not provided
- E72Q (p.Glu72Gln), NCI-TCGA Cosmic COSV5228, cosmic curated COSV52282, MetaLR 0.11, MetaSVM -0.99, Variant assessed as somatic; moderate impact.
- E75* (p.Glu75Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- E75K (p.Glu75Lys), cosmic curated COSV10499, TOPMed rs1431697220, gnomAD rs1431697220, REVEL 0.15, MetaLR 0.10, Uncertain significance, not provided; Inborn genetic diseases
- A77E (p.Ala77Glu), rs2510818969, ClinGen CA402244585, ClinVar RCV003127065, Uncertain significance, not provided
- A77T (p.Ala77Thr), rs767296927, ExAC rs767296927, gnomAD rs767296927, REVEL 0.05, MetaLR 0.07, Uncertain significance, not provided
- D78H (p.Asp78His), ExAC rs763887861, TOPMed rs763887861, gnomAD rs763887861
- D78N (p.Asp78Asn), ExAC rs763887861, TOPMed rs763887861, gnomAD rs763887861, REVEL 0.19, MetaLR 0.20
- D78Y (p.Asp78Tyr), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99296, Variant assessed as somatic; moderate impact.
- V81M (p.Val81Met), cosmic curated COSV10958, TOPMed rs1237757504
- D82E (p.Asp82Glu), ExAC rs762655258, gnomAD rs762655258
- E83G (p.Glu83Gly), ESP rs376492579, ExAC rs376492579, TOPMed rs376492579, gnomAD rs376492579, MetaLR 0.23, MetaSVM -0.82, Uncertain significance, Inborn genetic diseases
- E83K (p.Glu83Lys), cosmic curated COSV10586, NCI-TCGA TCGA novel, REVEL 0.16, MetaLR 0.15, Variant assessed as somatic; moderate impact.
- D84E (p.Asp84Glu), rs2144038346, ClinGen CA402244462, ClinVar RCV001979437, ClinVar RCV004044570, REVEL 0.46, MetaLR 0.31, Uncertain significance, Inborn genetic diseases; not provided
- D84G (p.Asp84Gly), rs373421991, ClinGen CA8923742, ClinVar RCV003842024, ESP rs373421991, REVEL 0.46, MetaLR 0.35, Uncertain significance, not provided
- G85D (p.Gly85Asp), NCI-TCGA Cosmic COSV5229, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99296, Variant assessed as somatic; moderate impact.
- G85V (p.Gly85Val), NCI-TCGA Cosmic COSV5229, cosmic curated COSV52298, NCI-TCGA Cosmic COSV9929, MetaLR 0.85, MetaSVM 0.87, Variant assessed as somatic; moderate impact.
- M86T (p.Met86Thr), ExAC rs773237462, gnomAD rs773237462, MetaLR 0.04, MetaSVM -1.06
- V87M (p.Val87Met), rs2510818892, ClinGen CA402244415, ClinVar RCV002303400, Uncertain significance, not provided
- A89V (p.Ala89Val), Ensembl rs868620601, MetaLR 0.23, MetaSVM -0.85
- V90L (p.Val90Leu), rs778990479, ClinGen CA8923738, ClinVar RCV002909630, ClinVar RCV002932314, REVEL 0.04, MetaLR 0.04, Uncertain significance, not provided; Inborn genetic diseases
- V90M (p.Val90Met), rs778990479, ClinGen CA8923737, cosmic curated COSV52290, ClinVar RCV001987001, REVEL 0.07, MetaLR 0.07, Uncertain significance, Inborn genetic diseases; not provided
- R91G (p.Arg91Gly), rs2510818861, ClinGen CA402244362, ClinVar RCV003301967, Uncertain significance, Inborn genetic diseases
- R91I (p.Arg91Ile), NCI-TCGA Cosmic COSV5227, cosmic curated COSV52279, MetaLR 0.34, MetaSVM -0.37, Variant assessed as somatic; moderate impact.
- S92G (p.Ser92Gly), rs150017015, ClinGen CA8923736, ClinVar RCV002141507, ClinVar RCV003903424, REVEL 0.07, MetaLR 0.08, Likely benign, not provided
- S92R (p.Ser92Arg), 1000Genomes rs150017015, ESP rs150017015, ExAC rs150017015, TOPMed rs150017015, REVEL 0.23, MetaLR 0.07, Conflicting interpretations, Inborn genetic diseases; not provided; Arrhythmogenic right ventricular cardiomy
- F93L (p.Phe93Leu), Ensembl rs2144038244, MetaLR 0.05, MetaSVM -1.07
- P94L (p.Pro94Leu), rs756638795, ClinGen CA8923733, ClinVar RCV002028480, ClinVar RCV005804461, REVEL 0.13, MetaLR 0.08, Uncertain significance, not provided; Inborn genetic diseases
- P94S (p.Pro94Ser), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99295, REVEL 0.07, MetaLR 0.11, Variant assessed as somatic; moderate impact.
- L95V (p.Leu95Val), TOPMed rs1354225874, Uncertain significance, Inborn genetic diseases
- S96F (p.Ser96Phe), NCI-TCGA TCGA novel, gnomAD rs1361176600, REVEL 0.17, MetaLR 0.30, Variant assessed as somatic; high impact.
- S97T (p.Ser97Thr), Ensembl rs2144038196, Uncertain significance, Inborn genetic diseases
- H99R (p.His99Arg), rs113785794, ClinGen CA8923731, ClinVar RCV002644086, ClinVar RCV005537540, REVEL 0.09, MetaLR 0.06, Conflicting interpretations, Inborn genetic diseases; not provided
- H99Y (p.His99Tyr), rs562222525, ClinGen CA8923732, ClinVar RCV003171565, ExAC rs562222525, REVEL 0.10, MetaLR 0.12, Likely benign, Inborn genetic diseases
- A100D (p.Ala100Asp), NCI-TCGA TCGA novel, MetaLR 0.27, MetaSVM -0.65, Variant assessed as somatic; moderate impact.
- K101M (p.Lys101Met), NCI-TCGA TCGA novel, MetaLR 0.09, MetaSVM -0.88, Variant assessed as somatic; moderate impact.
- K101N (p.Lys101Asn), TOPMed rs1404361272, REVEL 0.04, MetaLR 0.07
- K101R (p.Lys101Arg), gnomAD rs750207054, REVEL 0.06, MetaLR 0.06
- F102S (p.Phe102Ser), NCI-TCGA Cosmic COSV5229, cosmic curated COSV52292, MetaLR 0.43, MetaSVM -0.09, Variant assessed as somatic; moderate impact.
- L103V (p.Leu103Val), TOPMed rs1274222569, gnomAD rs1274222569, REVEL 0.07, MetaLR 0.06
- I104T (p.Ile104Thr), gnomAD rs1177369468, REVEL 0.34, MetaLR 0.15
- A106T (p.Ala106Thr), cosmic curated COSV52272, gnomAD rs1469377111, REVEL 0.60, MetaLR 0.58
- A106V (p.Ala106Val), rs2013164007, ClinGen CA402244258, ClinVar RCV003314193, Ensembl rs2013164007, REVEL 0.69, MetaLR 0.59, Uncertain significance, not provided
- Q107E (p.Gln107Glu), rs756870194, ClinGen CA8923730, ClinVar RCV003858663, ExAC rs756870194, REVEL 0.08, MetaLR 0.11, Uncertain significance, not provided
- D108Y (p.Asp108Tyr), ExAC rs751296292, gnomAD rs751296292, REVEL 0.83, MetaLR 0.68
- K109R (p.Lys109Arg), gnomAD rs1429699775, REVEL 0.05, MetaLR 0.05
- E110A (p.Glu110Ala), NCI-TCGA Cosmic COSV5227, cosmic curated COSV52272, MetaLR 0.14, MetaSVM -0.98, Variant assessed as somatic; moderate impact.
- E110Q (p.Glu110Gln), cosmic curated COSV99296, ExAC rs552668002, TOPMed rs552668002, gnomAD rs552668002, REVEL 0.14, MetaLR 0.14, Uncertain significance, not provided
- T111N (p.Thr111Asn), ExAC rs762857696
- T111S (p.Thr111Ser), rs2144038076, ClinGen CA402244226, ClinVar RCV001757500, Ensembl rs2144038076, AlphaMissense 0.10, MetaLR 0.09, Uncertain significance, not provided
- Q112P (p.Gln112Pro), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, Variant assessed as somatic; moderate impact.
- Q112R (p.Gln112Arg), rs368957587, ClinGen CA8923725, ClinVar RCV002321049, ClinVar RCV005058296, REVEL 0.08, MetaLR 0.09, Uncertain significance, not provided; Inborn genetic diseases
- W115* (p.Trp115Ter), rs2510818669, ClinGen CA402244194, ClinVar RCV003152213, CADD 38.00, Likely pathogenic
- W115L (p.Trp115Leu), NCI-TCGA TCGA novel, MetaLR 0.17, MetaSVM -0.93, Variant assessed as somatic; moderate impact.
- Q116* (p.Gln116Ter), gnomAD rs2013162892, CADD 41.00
- Q116L (p.Gln116Leu), NCI-TCGA Cosmic COSV5227, cosmic curated COSV52272, MetaLR 0.11, MetaSVM -0.92, Variant assessed as somatic; moderate impact.
- A118S (p.Ala118Ser), 1000Genomes rs17445840, ESP rs17445840, ExAC rs17445840, TOPMed rs17445840, MetaLR 0.08, MetaSVM -1.03, Benign
- A118T (p.Ala118Thr), rs17445840, ClinGen CA8923722, cosmic curated COSV52279, ClinVar RCV001681930, REVEL 0.03, MetaLR 0.01, Benign/Likely benign, not provided; not specified
- L121F (p.Leu121Phe), ExAC rs374765506, gnomAD rs374765506, REVEL 0.18, MetaLR 0.16, Uncertain significance, Inborn genetic diseases
- S122I (p.Ser122Ile), rs2510818624, ClinGen CA402244147, ClinVar RCV002840807, Uncertain significance, Inborn genetic diseases
- S122N (p.Ser122Asn), NCI-TCGA TCGA novel, MetaLR 0.12, MetaSVM -1.00, Variant assessed as somatic; moderate impact.
- L123P (p.Leu123Pro), rs2510818619, ClinGen CA402244141, ClinVar RCV003315070, Uncertain significance, not provided
- K124T (p.Lys124Thr), ExAC rs749692083, gnomAD rs749692083, MetaLR 0.10, MetaSVM -1.05
- T126I (p.Thr126Ile), rs770426519, ClinGen CA8923716, ClinVar RCV002009463, ClinVar RCV004046211, REVEL 0.09, AlphaMissense 0.07, Uncertain significance, Inborn genetic diseases; not provided
- T126N (p.Thr126Asn), rs770426519, ClinGen CA402244123, ClinVar RCV003288536, AlphaMissense 0.07, MetaLR 0.17, Uncertain significance, Inborn genetic diseases
- L127* (p.Leu127Ter), TOPMed rs1197514285
- L127F (p.Leu127Phe), rs971731737, ClinGen CA297918373, cosmic curated COSV52278, ClinVar RCV002927104, REVEL 0.04, MetaLR 0.10, Uncertain significance, Inborn genetic diseases; not provided
- L127V (p.Leu127Val), ExAC rs781533778, TOPMed rs781533778, gnomAD rs781533778, REVEL 0.05, MetaLR 0.09, Likely benign
- T128A (p.Thr128Ala), ExAC rs751016097, TOPMed rs751016097, gnomAD rs751016097, REVEL 0.04, MetaLR 0.09, Uncertain significance, not provided; Inborn genetic diseases
- T128I (p.Thr128Ile), ESP rs199902980, ExAC rs199902980, TOPMed rs199902980, gnomAD rs199902980, REVEL 0.04, MetaLR 0.12, Uncertain significance, not provided; Inborn genetic diseases
- T128P (p.Thr128Pro), ExAC rs751016097, TOPMed rs751016097, gnomAD rs751016097
- T128S (p.Thr128Ser), ExAC rs751016097, TOPMed rs751016097, gnomAD rs751016097, REVEL 0.04, MetaLR 0.10, Uncertain significance, Inborn genetic diseases; not provided
- E129K (p.Glu129Lys), rs963079228, NCI-TCGA Cosmic COSV5229, cosmic curated COSV52291, TOPMed rs963079228, AlphaMissense 0.07, MetaLR 0.12, Variant assessed as somatic; moderate impact.
- E130G (p.Glu130Gly), rs2510818553, ClinGen CA402244102, ClinVar RCV002899699, REVEL 0.09, MetaLR 0.15, Uncertain significance, not provided
- E130K (p.Glu130Lys), TOPMed rs2013160687, REVEL 0.12, MetaLR 0.13
- S131L (p.Ser131Leu), rs202040611, ClinGen CA8923708, ClinVar RCV003171564, ClinVar RCV004736320, REVEL 0.07, MetaLR 0.12, Uncertain significance, not provided; Inborn genetic diseases
- S131P (p.Ser131Pro), rs183606230, ClinGen CA8923709, ClinVar RCV001923765, ClinVar RCV003375448, REVEL 0.04, MetaLR 0.11, Uncertain significance, Inborn genetic diseases; not provided
- V132M (p.Val132Met), ExAC rs759313084, gnomAD rs759313084
- K133N (p.Lys133Asn), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99295, MetaLR 0.12, MetaSVM -0.98, Variant assessed as somatic; moderate impact.
- K133R (p.Lys133Arg), TOPMed rs980711081, gnomAD rs980711081, REVEL 0.06, MetaLR 0.14
- E134Q (p.Glu134Gln), TOPMed rs2013114932, gnomAD rs2013114932, REVEL 0.11, MetaLR 0.14
- E134V (p.Glu134Val), rs202032913, ClinGen CA8923689, ClinVar RCV002027302, ClinVar RCV002352755, REVEL 0.21, MetaLR 0.15, Conflicting interpretations, Inborn genetic diseases; not provided
- A136S (p.Ala136Ser), NCI-TCGA TCGA novel, MetaLR 0.11, MetaSVM -1.04, Variant assessed as somatic; moderate impact.
- E137K (p.Glu137Lys), gnomAD rs1248902182, REVEL 0.06, MetaLR 0.10
- E137V (p.Glu137Val), rs1396498254, ClinGen CA402244048, ClinVar RCV003898919, ClinVar RCV005311099, REVEL 0.10, MetaLR 0.17, Uncertain significance, Inborn genetic diseases
- V138A (p.Val138Ala), TOPMed rs1393606084, gnomAD rs1393606084, Uncertain significance
- V138D (p.Val138Asp), rs1393606084, ClinGen CA402244038, ClinVar RCV003182043, ClinVar RCV005061024, REVEL 0.11, MetaLR 0.15, Uncertain significance, Inborn genetic diseases; not provided
- V138I (p.Val138Ile), Ensembl rs1306883724
- E139K (p.Glu139Lys), rs1393676210, ClinGen CA402244037, ClinVar RCV002255041, ClinVar RCV003308081, REVEL 0.13, MetaLR 0.13, Uncertain significance, Inborn genetic diseases; not provided
- E139Q (p.Glu139Gln), TOPMed rs1393676210, gnomAD rs1393676210, REVEL 0.07, MetaLR 0.12, Uncertain significance
- E140* (p.Glu140Ter), NCI-TCGA Cosmic COSV5227, cosmic curated COSV52272, Variant assessed as somatic; high impact.
Public CDH2 analysis runs
- CDH2 analysis run — CDH2 (1,342 variants) — completed 2026-08-19