SRD5A2 (P31213) variants and mutations
SRD5A2 (also known as P31213) is a human protein-coding gene encoding a 3-oxo-5-alpha-steroid 4-dehydrogenase 2 protein. It converts testosterone to the more potent androgen dihydrotestosterone in androgen-responsive tissues. Biallelic loss-of-function variants cause 5-alpha-reductase type 2 deficiency, leading to undervirilization of 46,XY individuals and often increased virilization at puberty. This analysis covers 631 SRD5A2 variants and mutations. Of these, 97% have computational variant effect predictions. Disease context includes 46,XY disorder of sex development due to 5-alpha-reductase 2 deficiency, androgenetic alopecia, and benign prostatic hyperplasia. Example SRD5A2 variants include M1T, Q2E, and Q2L.
Variant analysis overview
- Gene: SRD5A2
- Protein: P31213
- UniProt accession: P31213
- Organism: Homo sapiens
- Variants analyzed: 631
- Variant scope: all variants
- Completed: 2026-08-22
Variant and mutation evidence
- Variant composition: 382 unspecified-consequence records; 1 natural variant; 1 stop retained variant; 16 frameshift variants; 1 stop lost; 72 synonymous variants; 135 missense variants; 12 stop-gained variants; 3 splice-region variants; 2 in-frame deletions; 11 substitution
- Prediction scores: 611 variants have prediction scores (97% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: 46,XY disorder of sex development due to 5-alpha-reductase 2 deficiency, androgenetic alopecia, benign prostatic hyperplasia, prostate carcinoma, prostate cancer, hypotrichosis, alopecia, Micropenis, hypogonadism, prostate neoplasm, neoplasm, lower urinary tract symptom.
Protein structure and variant hotspots
- Protein features: 4 transmembrane segments.
- Structural context: 179 variants have structural context.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable SRD5A2 variants
Examples include M1T, Q2E, Q2L, V3A, V3I, V3L, Q4*, Q4H. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1T (p.Met1Thr), rs886039748, ClinGen CA10588340, ClinVar RCV000254818, Pathogenic, not provided
- Q2E (p.Gln2Glu), gnomAD rs948700384, CADD 0.14, PolyPhen-2 0.03
- Q2L (p.Gln2Leu), NCI-TCGA Cosmic COSV5187, SIFT 0.43, Variant assessed as somatic; moderate impact.
- V3A (p.Val3Ala), ExAC rs755580189, gnomAD rs755580189, CADD 7.04, PolyPhen-2 0.01
- V3I (p.Val3Ile), ExAC rs763681675, TOPMed rs763681675, gnomAD rs763681675, CADD 0.57, PolyPhen-2 0.01, Uncertain significance, not specified
- V3L (p.Val3Leu), ExAC rs763681675, TOPMed rs763681675, gnomAD rs763681675, CADD 0.78, PolyPhen-2 0.01
- Q4* (p.Gln4Ter), rs2465708830, ClinGen CA346599293, ClinVar RCV002465022, Pathogenic
- Q4H (p.Gln4His), NCI-TCGA Cosmic COSV5187, Variant assessed as somatic; moderate impact.
- C5R (p.Cys5Arg), rs61748120, ClinGen CA224879, ClinVar RCV000083637, UniProt VAR 077546, AlphaMissense 0.82, not provided
- Q6* (p.Gln6Ter), rs9332960, ClinGen CA1600043, ClinVar RCV000500379, ClinVar RCV000578706, CADD 36.00, Pathogenic
- Q6X, rs9332960, Pathogenic
- Q7* (p.Gln7Ter), rs566562286, ClinGen CA346599272, ClinVar RCV003608508, 1000Genomes rs566562286, CADD 34.00, Pathogenic
- Q7E (p.Gln7Glu), 1000Genomes rs566562286, ExAC rs566562286, TOPMed rs566562286, gnomAD rs566562286, CADD 8.14, SIFT 1.00, Pathogenic
- P9A (p.Pro9Ala), NCI-TCGA Cosmic COSV9925, Variant assessed as somatic; moderate impact.
- P9S (p.Pro9Ser), rs868322910, ClinGen CA45142066, ClinVar RCV002006403, TOPMed rs868322910, CADD 13.90, PolyPhen-2 0.05, Uncertain significance, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- V10M (p.Val10Met), Ensembl rs1667068321, CADD 24.70, PolyPhen-2 1.00
- L11Q (p.Leu11Gln), ExAC rs759544280, TOPMed rs759544280, gnomAD rs759544280, CADD 24.20, PolyPhen-2 0.98
- A12E (p.Ala12Glu), rs2465708766, ClinGen CA346599240, ClinVar RCV003445401, CADD 23.80, PolyPhen-2 0.98, Likely pathogenic, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- G13D (p.Gly13Asp), ESP rs368219567, ExAC rs368219567, TOPMed rs368219567, gnomAD rs368219567, CADD 23.10, PolyPhen-2 1.00
- G13R (p.Gly13Arg), Ensembl rs1667068129, CADD 23.20, PolyPhen-2 1.00
- S14R (p.Ser14Arg), ExAC rs766177308, gnomAD rs766177308, CADD 24.40, PolyPhen-2 1.00
- A15D (p.Ala15Asp), TOPMed rs1468771535, SIFT 0.20
- A15T (p.Ala15Thr), NCI-TCGA Cosmic COSV5187, CADD 18.60, PolyPhen-2 0.06, Variant assessed as somatic; moderate impact.
- T16S (p.Thr16Ser), ExAC rs762683678, TOPMed rs762683678, gnomAD rs762683678, CADD 5.96, PolyPhen-2 0.01
- L17F (p.Leu17Phe), gnomAD rs1175535089, CADD 16.20, PolyPhen-2 0.90
- L17S (p.Leu17Ser), gnomAD rs1667067737, CADD 23.70, PolyPhen-2 0.95
- L17V (p.Leu17Val), gnomAD rs1405785453, CADD 16.70, PolyPhen-2 0.73
- V18I (p.Val18Ile), rs1457389420, TOPMed rs1457389420, gnomAD rs1457389420, CADD 3.27, PolyPhen-2 0.00, Variant assessed as somatic; moderate impact.
- A19T (p.Ala19Thr), NCI-TCGA Cosmic COSV5187, CADD 8.24, PolyPhen-2 0.01, Variant assessed as somatic; moderate impact.
- L20P (p.Leu20Pro), rs761824859, ClinGen CA1600035, ClinVar RCV000583658, ClinVar RCV001591351, CADD 23.00, PolyPhen-2 0.93, Pathogenic, not provided; 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- L20R (p.Leu20Arg), NCI-TCGA Cosmic COSV9925, CADD 22.80, PolyPhen-2 0.83, Variant assessed as somatic; moderate impact.
- L20V (p.Leu20Val), gnomAD rs1215794037, CADD 0.42, PolyPhen-2 0.22
- G21R (p.Gly21Arg), rs1265216982, gnomAD rs1265216982, ClinGen CA346599190, ClinVar RCV001940814, CADD 23.10, PolyPhen-2 1.00, Uncertain significance, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- A22S (p.Ala22Ser), gnomAD rs1217041314, CADD 6.62, PolyPhen-2 0.08
- A24V (p.Ala24Val), TOPMed rs1238726102, gnomAD rs1238726102, CADD 0.16, PolyPhen-2 0.00
- L25S (p.Leu25Ser), Ensembl rs1572375117
- Y26H (p.Tyr26His), gnomAD rs1305084717, CADD 15.70, PolyPhen-2 0.85
- A28E (p.Ala28Glu), ExAC rs781872598, CADD 0.99, PolyPhen-2 0.26
- A28T (p.Ala28Thr), ESP rs375737257, ExAC rs375737257, TOPMed rs375737257, gnomAD rs375737257, CADD 3.83, PolyPhen-2 0.02
- K29R (p.Lys29Arg), TOPMed rs1402454683, gnomAD rs1402454683, CADD 13.80, SIFT 0.66
- P30L (p.Pro30Leu), UniProt VAR 077547, CADD 23.40, PolyPhen-2 1.00, Uncertain significance
- S31C (p.Ser31Cys), ExAC rs782496734, TOPMed rs782496734, gnomAD rs782496734, CADD 18.40, PolyPhen-2 0.75, Benign
- S31F (p.Ser31Phe), rs782496734, ClinGen CA346599123, ClinVar RCV003608282, ExAC rs782496734, CADD 8.91, PolyPhen-2 0.03, Benign, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- S31P (p.Ser31Pro), Ensembl rs201096302
- G32S (p.Gly32Ser), rs781783385, ClinGen CA346599122, ClinVar RCV003501544, ExAC rs781783385, CADD 0.03, PolyPhen-2 0.01, Benign, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- G32V (p.Gly32Val), rs1328422263, ClinGen CA346599117, ClinVar RCV001511581, TOPMed rs1328422263, CADD 9.64, PolyPhen-2 0.26, Benign, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- G34R (p.Gly34Arg), rs782032018, ClinGen CA346599107, ClinVar RCV001030762, UniProt VAR 087981, CADD 25.60, PolyPhen-2 1.00, Pathogenic, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- K35N (p.Lys35Asn), ExAC rs782766740, TOPMed rs782766740
- K35Q (p.Lys35Gln), Ensembl rs1667065974, SIFT 0.00
- H36Q (p.His36Gln), gnomAD rs1487065913, CADD 16.70, PolyPhen-2 0.03
- H36R (p.His36Arg), TOPMed rs1187445751, gnomAD rs1187445751, CADD 23.30, PolyPhen-2 0.46
- T37A (p.Thr37Ala), ExAC rs782140524, TOPMed rs782140524, gnomAD rs782140524, CADD 0.20, PolyPhen-2 0.00, Uncertain significance, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- T37P (p.Thr37Pro), ExAC rs782140524, TOPMed rs782140524, gnomAD rs782140524, CADD 3.66, PolyPhen-2 0.16
- T37R (p.Thr37Arg), NCI-TCGA TCGA novel, CADD 0.18, PolyPhen-2 0.21, Variant assessed as somatic; moderate impact.
- E38* (p.Glu38Ter), TOPMed rs1347898502, gnomAD rs1347898502, CADD 32.00
- E38A (p.Glu38Ala), ExAC rs761623469, gnomAD rs761623469, CADD 9.95, PolyPhen-2 0.03
- E38G (p.Glu38Gly), ExAC rs761623469, gnomAD rs761623469, SIFT 0.38
- E38K (p.Glu38Lys), TOPMed rs1347898502, gnomAD rs1347898502, CADD 3.50, PolyPhen-2 0.03
- P42A (p.Pro42Ala), ExAC rs762742772, gnomAD rs762742772, CADD 6.38, PolyPhen-2 0.29
- P42L (p.Pro42Leu), NCI-TCGA Cosmic COSV9925, CADD 20.30, PolyPhen-2 0.68, Variant assessed as somatic; moderate impact.
- P42Q (p.Pro42Gln), ExAC rs750200112, gnomAD rs750200112, CADD 15.50, PolyPhen-2 0.31
- P42S (p.Pro42Ser), NCI-TCGA Cosmic COSV9925, SIFT 0.19, Variant assessed as somatic; moderate impact.
- A43V (p.Ala43Val), TOPMed rs1667065160, CADD 0.68, PolyPhen-2 0.00
- A44T (p.Ala44Thr), rs1435250396, gnomAD rs1435250396, CADD 6.31, PolyPhen-2 0.03, Variant assessed as somatic; moderate impact.
- A44V (p.Ala44Val), ExAC rs765140743, TOPMed rs765140743, gnomAD rs765140743, CADD 3.08, PolyPhen-2 0.01
- T45A (p.Thr45Ala), ExAC rs762020997, gnomAD rs762020997, CADD 0.02, PolyPhen-2 0.00
- T45I (p.Thr45Ile), ExAC rs776884291, TOPMed rs776884291, gnomAD rs776884291, CADD 2.58, PolyPhen-2 0.00
- T45N (p.Thr45Asn), ExAC rs776884291, TOPMed rs776884291, gnomAD rs776884291, CADD 2.01, PolyPhen-2 0.09
- T45S (p.Thr45Ser), ExAC rs776884291, TOPMed rs776884291, gnomAD rs776884291, CADD 1.24, PolyPhen-2 0.01
- R46C (p.Arg46Cys), rs914715976, NCI-TCGA Cosmic COSV5187, TOPMed rs914715976, CADD 2.86, PolyPhen-2 0.01, Variant assessed as somatic; moderate impact.
- R46G (p.Arg46Gly), TOPMed rs914715976
- R46H (p.Arg46His), ExAC rs768670705, TOPMed rs768670705, gnomAD rs768670705, CADD 11.10, PolyPhen-2 0.01
- R46L (p.Arg46Leu), ExAC rs768670705, TOPMed rs768670705, gnomAD rs768670705, CADD 8.86, PolyPhen-2 0.01
- L47M (p.Leu47Met), TOPMed rs1215174536
- P48L (p.Pro48Leu), rs61748122, ClinGen CA1600024, ClinVar RCV000695133, ExAC rs61748122, CADD 24.90, PolyPhen-2 0.91, Uncertain significance, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- P48R (p.Pro48Arg), rs61748122, ClinGen CA224882, ClinVar RCV000083639, UniProt VAR 077548, CADD 24.50, PolyPhen-2 0.93, not provided
- P48T (p.Pro48Thr), TOPMed rs1260097640, gnomAD rs1260097640, CADD 20.80, PolyPhen-2 0.83
- A49D (p.Ala49Asp), ESP rs370278229, ExAC rs370278229, TOPMed rs370278229, gnomAD rs370278229, CADD 24.40, PolyPhen-2 0.84
- A49T (p.Ala49Thr), rs9282858, ClinGen CA116154, ClinVar RCV000003511, ClinVar RCV000083640, CADD 20.90, PolyPhen-2 0.38, Benign, not provided; 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- A49V (p.Ala49Val), ESP rs370278229, ExAC rs370278229, TOPMed rs370278229, gnomAD rs370278229, CADD 24.20, PolyPhen-2 0.78
- R50G (p.Arg50Gly), rs369117426, NCI-TCGA Cosmic COSV5187, ESP rs369117426, ExAC rs369117426, CADD 21.20, PolyPhen-2 0.01, Variant assessed as somatic; moderate impact.
- R50H (p.Arg50His), rs372049682, NCI-TCGA Cosmic COSV5187, ExAC rs372049682, TOPMed rs372049682, CADD 23.50, PolyPhen-2 0.83, Variant assessed as somatic; moderate impact.
- R50S (p.Arg50Ser), ESP rs369117426, ExAC rs369117426, TOPMed rs369117426, gnomAD rs369117426, CADD 20.90, PolyPhen-2 0.07
- A51S (p.Ala51Ser), ExAC rs61748123, TOPMed rs61748123, gnomAD rs61748123, CADD 15.20, PolyPhen-2 0.61, Uncertain significance
- A51T (p.Ala51Thr), rs61748123, ClinGen CA224884, ClinVar RCV000083641, ClinVar RCV004767064, CADD 10.10, PolyPhen-2 0.08, Conflicting interpretations, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- A52S (p.Ala52Ser), 1000Genomes rs564403641, ExAC rs564403641, TOPMed rs564403641, gnomAD rs564403641, CADD 24.00, PolyPhen-2 0.93, Likely pathogenic
- A52T (p.Ala52Thr), rs564403641, ClinGen CA1600019, NCI-TCGA Cosmic COSV5187, ClinVar RCV001576730, CADD 24.60, PolyPhen-2 0.97, Likely pathogenic, not provided
- W53* (p.Trp53Ter), rs1667063572, ClinGen CA346599001, ClinVar RCV003501687, gnomAD rs1667063572, CADD 37.00, Pathogenic
- L55M (p.Leu55Met), NCI-TCGA Cosmic COSV9925, CADD 23.30, PolyPhen-2 0.95, Variant assessed as somatic; moderate impact., in PPSH
- L55P (p.Leu55Pro), rs121434245, ClinGen CA346598986, ClinVar RCV001270011, ClinVar RCV002272440, CADD 26.20, PolyPhen-2 0.97, Pathogenic/Likely pathogenic, not provided; 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- L55Q (p.Leu55Gln), rs121434245, ClinGen CA340068, ClinVar RCV000003503, ClinVar RCV001269601, CADD 25.00, PolyPhen-2 0.48, Pathogenic/Likely pathogenic, not provided; Urogenital tract malformation; 3-Oxo-5 alpha-steroid delta 4-dehyd
- Q56* (p.Gln56Ter), Ensembl rs1667063250, CADD 37.00
- Q56H (p.Gln56His), gnomAD rs1311014616, CADD 21.40, PolyPhen-2 0.99
- Q56K (p.Gln56Lys), NCI-TCGA Cosmic COSV9925, CADD 24.40, PolyPhen-2 0.89, Variant assessed as somatic; moderate impact.
- Q56R (p.Gln56Arg), rs1357268588, ClinGen CA346598980, ClinVar RCV003501686, ClinVar RCV004701727, CADD 24.40, PolyPhen-2 0.62, Conflicting interpretations, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency; not specified
- E57* (p.Glu57Ter), rs750444774, ClinGen CA346598976, ClinVar RCV001726692, ClinVar RCV001726693, AlphaMissense 0.87, Pathogenic
- E57A (p.Glu57Ala), TOPMed rs1401586494, gnomAD rs1401586494, SIFT 0.00
- E57Q (p.Glu57Gln), rs750444774, ClinGen CA1600017, ClinVar RCV000582093, ExAC rs750444774, AlphaMissense 0.87, CADD 24.20, Pathogenic, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- P59L (p.Pro59Leu), gnomAD rs1009792956, CADD 26.00, PolyPhen-2 1.00
- F61L (p.Phe61Leu), TOPMed rs61750385, gnomAD rs61750385, CADD 10.40, PolyPhen-2 0.22, Likely benign
- A62S (p.Ala62Ser), TOPMed rs1340733222, gnomAD rs1340733222, CADD 17.50, PolyPhen-2 0.47
- A62T (p.Ala62Thr), NCI-TCGA Cosmic COSV5187, TOPMed rs1340733222, gnomAD rs1340733222, CADD 15.40, PolyPhen-2 0.21, Variant assessed as somatic; moderate impact.
- A62V (p.Ala62Val), NCI-TCGA Cosmic COSV5187, Ensembl rs1572374876, CADD 1.21, PolyPhen-2 0.00, Variant assessed as somatic; moderate impact.
- V63M (p.Val63Met), gnomAD rs1475766670
- P64L (p.Pro64Leu), rs2465708311, ClinGen CA346598928, ClinVar RCV002968585, CADD 25.30, PolyPhen-2 0.91, Uncertain significance, Inborn genetic diseases
- A65P (p.Ala65Pro), rs1186430097, ClinGen CA346598926, ClinVar RCV001269740, ClinVar RCV003500674, CADD 22.70, PolyPhen-2 0.94, Pathogenic/Likely pathogenic, not provided; 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- A65S (p.Ala65Ser), TOPMed rs1186430097, gnomAD rs1186430097, SIFT 0.20, Pathogenic
- A65T (p.Ala65Thr), rs1186430097, NCI-TCGA Cosmic COSV5187, TOPMed rs1186430097, gnomAD rs1186430097, CADD 14.60, PolyPhen-2 0.18, Pathogenic, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- A65V (p.Ala65Val), TOPMed rs1667061819, CADD 4.08, PolyPhen-2 0.03
- G66E (p.Gly66Glu), NCI-TCGA Cosmic COSV5187, Variant assessed as somatic; moderate impact.
- G66R (p.Gly66Arg), rs550866120, ClinGen CA1600013, ClinVar RCV003317732, ClinVar RCV003777292, CADD 22.20, PolyPhen-2 0.92, Conflicting interpretations, not specified; 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- G66V (p.Gly66Val), gnomAD rs1250601374, CADD 12.00, PolyPhen-2 0.28
- I67F (p.Ile67Phe), ESP rs371573955, ExAC rs371573955, TOPMed rs371573955, gnomAD rs371573955, CADD 14.20, PolyPhen-2 0.03
- I67S (p.Ile67Ser), ESP rs376673386, TOPMed rs376673386, gnomAD rs376673386, CADD 23.20, PolyPhen-2 0.64
- L68F (p.Leu68Phe), TOPMed rs1233627532, gnomAD rs1233627532, CADD 23.00, PolyPhen-2 0.39
- L68I (p.Leu68Ile), NCI-TCGA TCGA novel, CADD 20.80, PolyPhen-2 0.40, Variant assessed as somatic; moderate impact.
- L68V (p.Leu68Val), TOPMed rs1233627532, gnomAD rs1233627532, CADD 22.90, PolyPhen-2 0.75
- A69S (p.Ala69Ser), rs1553329443, ClinGen CA346598903, ClinVar RCV000583779, Ensembl rs1553329443, CADD 18.20, PolyPhen-2 0.61, Pathogenic, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- A69T (p.Ala69Thr), NCI-TCGA Cosmic COSV9925, CADD 14.90, PolyPhen-2 0.08, Variant assessed as somatic; moderate impact.
- R70Q (p.Arg70Gln), rs61750387, ClinGen CA224893, ClinVar RCV000083646, TOPMed rs61750387, CADD 2.87, PolyPhen-2 0.01, not provided
- R70W (p.Arg70Trp), ExAC rs771374873, TOPMed rs771374873, gnomAD rs771374873, CADD 15.00, PolyPhen-2 0.00
- Q71* (p.Gln71Ter), rs1060499834, ClinGen CA16609845, ClinVar RCV000469192, TOPMed rs1060499834, CADD 36.00, Pathogenic
- P72L (p.Pro72Leu), TOPMed rs1393252721, gnomAD rs1393252721, CADD 22.00, PolyPhen-2 0.25
- P72R (p.Pro72Arg), TOPMed rs1393252721, gnomAD rs1393252721, SIFT 0.18
- P72S (p.Pro72Ser), rs61748124, ClinGen CA224897, ClinVar RCV000083648, Ensembl rs61748124, CADD 10.20, PolyPhen-2 0.02, not provided
- L73F (p.Leu73Phe), TOPMed rs1398349933, gnomAD rs1398349933, CADD 12.30, PolyPhen-2 0.06
- L73I (p.Leu73Ile), TOPMed rs1398349933, gnomAD rs1398349933, CADD 10.20, PolyPhen-2 0.00
- L73P (p.Leu73Pro), Ensembl rs1667057376, CADD 7.08, PolyPhen-2 0.00
- S74C (p.Ser74Cys), TOPMed rs1462234672, gnomAD rs1462234672, CADD 14.10, PolyPhen-2 0.02
- S74F (p.Ser74Phe), TOPMed rs1462234672, gnomAD rs1462234672, CADD 14.50, PolyPhen-2 0.01
- L75F (p.Leu75Phe), TOPMed rs1422094082, gnomAD rs1422094082, CADD 11.10, SIFT 0.16
- G77E (p.Gly77Glu), rs886055955, ClinGen CA10613215, ClinVar RCV002519968, Ensembl rs886055955, CADD 13.30, PolyPhen-2 0.12, Uncertain significance, Inborn genetic diseases
- G77R (p.Gly77Arg), ExAC rs746737164, gnomAD rs746737164, CADD 11.20, PolyPhen-2 0.05
- P78A (p.Pro78Ala), TOPMed rs763591035
- P78T (p.Pro78Thr), TOPMed rs763591035, CADD 12.00, PolyPhen-2 0.01
- P79S (p.Pro79Ser), TOPMed rs1237144251, gnomAD rs1237144251, CADD 21.10, PolyPhen-2 0.23
- P79T (p.Pro79Thr), TOPMed rs1237144251, gnomAD rs1237144251, CADD 22.70, PolyPhen-2 0.23
- G80W (p.Gly80Trp), gnomAD rs1304538007, CADD 19.10, PolyPhen-2 0.03
- T81M (p.Thr81Met), Ensembl rs1667056569, CADD 14.60, PolyPhen-2 0.45
- L83R (p.Leu83Arg), NCI-TCGA Cosmic COSV5187, NCI-TCGA Cosmic COSV9925, Variant assessed as somatic; moderate impact.
- L84M (p.Leu84Met), 1000Genomes rs369626334, ESP rs369626334, ExAC rs369626334, TOPMed rs369626334, CADD 24.30, PolyPhen-2 0.96
- G85D (p.Gly85Asp), rs1351269392, UniProt VAR 013130, TOPMed rs1351269392, gnomAD rs1351269392, CADD 23.40, PolyPhen-2 0.66, Pathogenic, in PPSH
- G85S (p.Gly85Ser), ExAC rs778850680, gnomAD rs778850680, CADD 19.90, PolyPhen-2 0.25
- L86P (p.Leu86Pro), gnomAD rs1374773126, CADD 23.60, PolyPhen-2 0.04
- L86V (p.Leu86Val), ExAC rs756975134, gnomAD rs756975134, CADD 18.60, PolyPhen-2 0.08
- F87I (p.Phe87Ile), NCI-TCGA TCGA novel, SIFT 0.00, Variant assessed as somatic; moderate impact.
- C88F (p.Cys88Phe), TOPMed rs868416832, gnomAD rs868416832, CADD 23.30, PolyPhen-2 0.86
- C88W (p.Cys88Trp), TOPMed rs867198056, SIFT 0.05, Benign
- C88Y (p.Cys88Tyr), TOPMed rs868416832, gnomAD rs868416832, CADD 23.20, PolyPhen-2 0.93
- L89I (p.Leu89Ile), 1000Genomes rs523349, ESP rs523349, ExAC rs523349, TOPMed rs523349, CADD 5.44, PolyPhen-2 0.01, Benign
- L89P (p.Leu89Pro), gnomAD rs1321956713, CADD 14.90, PolyPhen-2 0.10
- L89V (p.Leu89Val), rs2465708158, ClinGen CA2740092818, ClinVar RCV003855105, CADD 1.52, PolyPhen-2 0.00, Likely benign, not specified; not provided; 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficie
- Y91C (p.Tyr91Cys), gnomAD rs1171940374, CADD 27.10, PolyPhen-2 0.97
- Y91D (p.Tyr91Asp), rs201175894, ClinGen CA1599995, ClinVar RCV000581450, ClinVar RCV004767421, CADD 24.30, PolyPhen-2 0.25, Uncertain significance, not specified
- Y91H (p.Tyr91His), rs201175894, ClinGen CA1599996, ClinVar RCV000582682, ClinVar RCV001821707, CADD 24.20, PolyPhen-2 0.25, Pathogenic/Likely pathogenic, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency; not provided
- Y91N (p.Tyr91Asn), ExAC rs201175894, TOPMed rs201175894, gnomAD rs201175894, CADD 27.00, SIFT 0.00, Pathogenic
- F92L (p.Phe92Leu), TOPMed rs895624262, gnomAD rs895624262, CADD 22.50, PolyPhen-2 0.47
- F92Y (p.Phe92Tyr), gnomAD rs1379165497, SIFT 0.03
- H93N (p.His93Asn), gnomAD rs1455300003, CADD 20.20, PolyPhen-2 0.03
- H93Y (p.His93Tyr), gnomAD rs1455300003, CADD 16.30, PolyPhen-2 0.01
- R94G (p.Arg94Gly), Ensembl rs1348710658, CADD 31.00, PolyPhen-2 0.96
- R94K (p.Arg94Lys), gnomAD rs1244660622, CADD 29.70, PolyPhen-2 0.89
- R94M (p.Arg94Met), rs867958346, []
- T95I (p.Thr95Ile), rs891598499, ClinGen CA45136786, ClinVar RCV003501148, TOPMed rs891598499, CADD 24.20, PolyPhen-2 0.99, Uncertain significance, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- F96L (p.Phe96Leu), 1000Genomes rs562449429, ExAC rs562449429, TOPMed rs562449429, gnomAD rs562449429, CADD 16.40, PolyPhen-2 0.52
- F96S (p.Phe96Ser), NCI-TCGA TCGA novel, CADD 25.10, PolyPhen-2 0.99, Variant assessed as somatic; moderate impact.
- V97L (p.Val97Leu), ExAC rs774936492, gnomAD rs774936492, CADD 16.50, PolyPhen-2 0.13
- L101F (p.Leu101Phe), ExAC rs201312221, gnomAD rs201312221, CADD 15.80, PolyPhen-2 0.03
- N102D (p.Asn102Asp), gnomAD rs1477387133, CADD 22.10, PolyPhen-2 0.04
- N102K (p.Asn102Lys), gnomAD rs1339954526, SIFT 0.15
- N102S (p.Asn102Ser), rs1418439291, NCI-TCGA Cosmic COSV5187, TOPMed rs1418439291, gnomAD rs1418439291, CADD 6.48, PolyPhen-2 0.00, Variant assessed as somatic; moderate impact.
- R103* (p.Arg103Ter), rs267599353, ClinGen CA1599969, ClinVar RCV000634579, ClinVar RCV001270012, CADD 35.00, SIFT 0.01, Pathogenic
- R103L (p.Arg103Leu), NCI-TCGA Cosmic COSV5187, NCI-TCGA Cosmic COSV9925, CADD 24.00, PolyPhen-2 0.99, Variant assessed as somatic; moderate impact.
- R103Q (p.Arg103Gln), rs749199514, NCI-TCGA Cosmic COSV5187, NCI-TCGA Cosmic COSV9925, ExAC rs749199514, CADD 22.90, PolyPhen-2 0.98, Variant assessed as somatic; moderate impact.
- G104E (p.Gly104Glu), rs777711528, ClinGen CA1599966, ClinVar RCV003459918, ExAC rs777711528, CADD 23.50, PolyPhen-2 0.99, Pathogenic, 3-Oxo-5 alpha-steroid delta 4-dehydrogenase deficiency
- G104R (p.Gly104Arg), TOPMed rs1443380453, CADD 23.70, PolyPhen-2 0.99
- G104W (p.Gly104Trp), TOPMed rs1443380453, CADD 24.30, PolyPhen-2 1.00
- R105K (p.Arg105Lys), 1000Genomes rs148028901, TOPMed rs148028901, gnomAD rs148028901, CADD 12.30, PolyPhen-2 0.23
- P106A (p.Pro106Ala), ExAC rs769436494, TOPMed rs769436494, gnomAD rs769436494, CADD 17.20, PolyPhen-2 0.21
- P106L (p.Pro106Leu), ExAC rs747979984, TOPMed rs747979984, gnomAD rs747979984, CADD 22.40, PolyPhen-2 0.30
Public SRD5A2 analysis runs
- SRD5A2 analysis run — SRD5A2 (631 variants) — completed 2026-08-22