ALDOB (Fructose-bisphosphate aldolase B) variants and mutations
ALDOB (also known as Fructose-bisphosphate aldolase B) is a human protein-coding gene encoding a fructose-bisphosphate aldolase B protein. It cleaves fructose-1-phosphate and fructose-1,6-bisphosphate during fructose and glucose metabolism in liver, kidney, and intestine. Biallelic loss-of-function variants cause hereditary fructose intolerance, in which fructose ingestion can trigger hypoglycemia, vomiting, and liver injury. This analysis covers 814 ALDOB variants and mutations. Of these, 79% have computational variant effect predictions. Disease context includes hereditary fructose intolerance, hereditary disease, and acute liver failure. Example ALDOB variants include M1L, M1R, and M1T.
Variant analysis overview
- Gene: ALDOB
- Protein: Fructose-bisphosphate aldolase B
- UniProt accession: P05062
- Organism: Homo sapiens
- Variants analyzed: 814
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 595 unspecified-consequence records; 106 missense variants; 89 synonymous variants; 5 in-frame deletions; 11 frameshift variants; 5 splice-region variants; 1 stop lost; 3 stop-gained variants; 1 in-frame insertions; 1 substitution
- Prediction scores: 640 variants have prediction scores (79% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: hereditary fructose intolerance, hereditary disease, acute liver failure, disorder of glycogen metabolism, carbohydrate metabolism disease, hepatocellular carcinoma, neoplasm, Genu valgum, Genu varum, nonpapillary renal cell carcinoma, gastric cancer, cancer.
Protein structure and variant hotspots
- Protein features: 3 binding sites; 14 post-translational modification sites.
- PTM context: 32 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable ALDOB variants
Examples include M1L, M1R, M1T, M1V, A2T, A2V, H3Q, R4*. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1L (p.Met1Leu), rs2490130765, ClinGen CA374266323, ClinVar RCV003599815, Likely pathogenic, Hereditary fructosuria
- M1R (p.Met1Arg), rs1270747182, ClinGen CA374266320, ClinVar RCV003048085, MetaLR 0.80, MetaSVM 0.75, Likely pathogenic, Hereditary fructosuria
- M1T (p.Met1Thr), rs1270747182, ClinGen CA374266321, ClinVar RCV001215627, MetaLR 0.80, MetaSVM 0.75, Pathogenic/Likely pathogenic, Hereditary fructosuria
- M1V (p.Met1Val), rs2490130765, ClinGen CA374266324, ClinVar RCV003084680, Likely pathogenic, Hereditary fructosuria
- A2T (p.Ala2Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A2V (p.Ala2Val), rs930944969, ClinGen CA196958401, ClinVar RCV002879403, TOPMed rs930944969, CADD 22.40, PolyPhen-2 0.10, Uncertain significance, Inborn genetic diseases
- H3Q (p.His3Gln), gnomAD rs1345378132, CADD 15.40, PolyPhen-2 0.01
- R4* (p.Arg4Ter), rs118204428, ClinGen CA114310, ClinVar RCV000000500, ExAC rs118204428, CADD 37.00, Pathogenic
- R4G (p.Arg4Gly), ExAC rs118204428, TOPMed rs118204428, gnomAD rs118204428, Pathogenic
- R4L (p.Arg4Leu), ExAC rs767812270, gnomAD rs767812270, CADD 14.80, PolyPhen-2 0.00
- R4P (p.Arg4Pro), ExAC rs767812270, gnomAD rs767812270, CADD 15.20
- R4Q (p.Arg4Gln), rs767812270, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, ExAC rs767812270, CADD 8.71, PolyPhen-2 0.00, Variant assessed as somatic; moderate impact.
- F5C (p.Phe5Cys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P6A (p.Pro6Ala), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, Variant assessed as somatic; moderate impact.
- P6L (p.Pro6Leu), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, Variant assessed as somatic; moderate impact.
- P6R (p.Pro6Arg), Ensembl rs2118366455, CADD 25.00, PolyPhen-2 0.95
- T9A (p.Thr9Ala), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 22.00, PolyPhen-2 0.01, Variant assessed as somatic; moderate impact.
- T9I (p.Thr9Ile), TOPMed rs1588172747, Uncertain significance, Inborn genetic diseases
- T9N (p.Thr9Asn), cosmic curated COSV10087, TOPMed rs1588172747, CADD 17.20, PolyPhen-2 0.02, Uncertain significance
- Q10H (p.Gln10His), ESP rs376852683, TOPMed rs376852683, gnomAD rs376852683, CADD 15.40
- Q10R (p.Gln10Arg), Ensembl rs1831209537
- E11D (p.Glu11Asp), 1000Genomes rs544090689, ExAC rs544090689, gnomAD rs544090689, CADD 7.51, PolyPhen-2 0.00, Uncertain significance, ALDOB-related disorder
- Q12* (p.Gln12Ter), rs190631679, ClinGen CA374266252, ClinVar RCV001941654, 1000Genomes rs190631679, CADD 36.00, Pathogenic
- Q12E (p.Gln12Glu), 1000Genomes rs190631679, Pathogenic
- K13N (p.Lys13Asn), ExAC rs751674905, gnomAD rs751674905, CADD 24.90, PolyPhen-2 0.81
- K13Q (p.Lys13Gln), rs2490130664, ClinGen CA374266246, ClinVar RCV003496836, Uncertain significance, Hereditary fructosuria
- K13R (p.Lys13Arg), NCI-TCGA Cosmic COSV6639, Variant assessed as somatic; moderate impact.
- K13T (p.Lys13Thr), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, Variant assessed as somatic; moderate impact.
- K14E (p.Lys14Glu), gnomAD rs1352286264, CADD 21.90, PolyPhen-2 0.00
- K14R (p.Lys14Arg), Ensembl rs891959617, CADD 22.70, PolyPhen-2 0.01
- L16F (p.Leu16Phe), ExAC rs761836485, gnomAD rs761836485, CADD 26.10, PolyPhen-2 1.00
- L16H (p.Leu16His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L16V (p.Leu16Val), ExAC rs761836485, gnomAD rs761836485
- S17L (p.Ser17Leu), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, TOPMed rs1755846651, Variant assessed as somatic; moderate impact.
- E18* (p.Glu18Ter), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, CADD 36.00, Variant assessed as somatic; high impact.
- E18D (p.Glu18Asp), TOPMed rs1407298203, gnomAD rs1407298203
- A20S (p.Ala20Ser), rs575202673, NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, 1000Genomes rs575202673, CADD 24.70, PolyPhen-2 0.96, Variant assessed as somatic; moderate impact.
- A20V (p.Ala20Val), ExAC rs763957973, TOPMed rs763957973, gnomAD rs763957973, CADD 24.10, PolyPhen-2 0.42
- Q21* (p.Gln21Ter), rs2118366288, ClinGen CA374266194, ClinVar RCV001920274, Ensembl rs2118366288, Pathogenic
- Q21E (p.Gln21Glu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- Q21H (p.Gln21His), cosmic curated COSV66398, Ensembl rs769234802, CADD 11.90, PolyPhen-2 0.00
- S22G (p.Ser22Gly), rs1831208641, ClinGen CA374266186, ClinVar RCV002702961, TOPMed rs1831208641, AlphaMissense 0.07, MetaLR 0.33, Uncertain significance, Inborn genetic diseases
- I23L (p.Ile23Leu), gnomAD rs1428910288, CADD 22.50, PolyPhen-2 0.23
- A25T (p.Ala25Thr), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, Uncertain significance, Hereditary fructosuria
- A25V (p.Ala25Val), cosmic curated COSV66397, TOPMed rs1178025343, gnomAD rs1178025343, CADD 23.60, PolyPhen-2 0.05, Uncertain significance, Hereditary fructosuria
- N26I (p.Asn26Ile), 1000Genomes rs186949752, ExAC rs186949752, TOPMed rs186949752, gnomAD rs186949752, CADD 23.50, PolyPhen-2 0.20
- N26K (p.Asn26Lys), cosmic curated COSV66398, gnomAD rs1180910257, CADD 22.20, PolyPhen-2 0.01, Likely benign
- N26S (p.Asn26Ser), 1000Genomes rs186949752, ExAC rs186949752, TOPMed rs186949752, gnomAD rs186949752, CADD 20.00, PolyPhen-2 0.00
- N26Y (p.Asn26Tyr), rs760539963, ClinGen CA5161750, ClinVar RCV003225854, ExAC rs760539963, CADD 23.00, PolyPhen-2 0.44, Uncertain significance, Hereditary fructosuria
- G27A (p.Gly27Ala), TOPMed rs1831208245, CADD 25.30, PolyPhen-2 0.99, Uncertain significance, Inborn genetic diseases
- K28N (p.Lys28Asn), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 25.20, PolyPhen-2 0.94, Variant assessed as somatic; moderate impact.
- K28T (p.Lys28Thr), TOPMed rs1198906346, gnomAD rs1198906346, CADD 27.10, PolyPhen-2 0.94
- G29E (p.Gly29Glu), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 25.90, PolyPhen-2 1.00, Variant assessed as somatic; moderate impact.
- G29R (p.Gly29Arg), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, gnomAD rs1264756715, CADD 26.50, PolyPhen-2 1.00, Uncertain significance, Hereditary fructosuria
- I30N (p.Ile30Asn), Ensembl rs781067490, CADD 28.60, PolyPhen-2 1.00
- L31M (p.Leu31Met), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, NCI-TCGA Cosmic COSV9905, Variant assessed as somatic; moderate impact.
- A32P (p.Ala32Pro), rs1831207922, ClinGen CA374266123, ClinVar RCV001167308, gnomAD rs1831207922, CADD 27.30, PolyPhen-2 1.00, Uncertain significance, Hereditary fructosuria
- A32T (p.Ala32Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A33V (p.Ala33Val), Ensembl rs1831207811, CADD 26.50, PolyPhen-2 0.95
- D34E (p.Asp34Glu), 1000Genomes rs181247220, ExAC rs181247220, gnomAD rs181247220, CADD 24.60, PolyPhen-2 0.97
- S36T (p.Ser36Thr), gnomAD rs1370456880, CADD 26.20, PolyPhen-2 0.76
- V37L (p.Val37Leu), TOPMed rs1278516998, gnomAD rs1278516998, CADD 22.90, PolyPhen-2 0.00
- T39A (p.Thr39Ala), gnomAD rs1317153259
- M40R (p.Met40Arg), ESP rs77849749, ExAC rs77849749, TOPMed rs77849749, gnomAD rs77849749
- M40T (p.Met40Thr), ESP rs77849749, ExAC rs77849749, TOPMed rs77849749, gnomAD rs77849749, CADD 23.50, PolyPhen-2 0.31
- M40V (p.Met40Val), TOPMed rs1831193453, CADD 21.40, PolyPhen-2 0.04
- G41R (p.Gly41Arg), ExAC rs755336557, TOPMed rs755336557, gnomAD rs755336557, CADD 26.00, PolyPhen-2 0.97, Uncertain significance, Inborn genetic diseases
- N42T (p.Asn42Thr), Ensembl rs1588172391, NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- R43C (p.Arg43Cys), rs772473508, ClinGen CA5161719, ClinVar RCV001167306, ClinVar RCV004590111, CADD 29.60, PolyPhen-2 0.99, Uncertain significance, not provided; Hereditary fructosuria
- R43H (p.Arg43His), rs780442649, ClinGen CA5161718, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, CADD 28.10, PolyPhen-2 0.95, Uncertain significance, not provided; Hereditary fructosuria
- R43L (p.Arg43Leu), rs780442649, ClinGen CA374266040, ClinVar RCV001771072, ExAC rs780442649, CADD 27.90, PolyPhen-2 1.00, Uncertain significance, not provided
- L44V (p.Leu44Val), TOPMed rs1387179219, gnomAD rs1387179219, CADD 25.30, PolyPhen-2 0.82
- Q45* (p.Gln45Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- Q45H (p.Gln45His), cosmic curated COSV10087, Ensembl rs1013015077, CADD 23.50, PolyPhen-2 0.61
- Q45R (p.Gln45Arg), ExAC rs758508874, gnomAD rs758508874, CADD 22.20, PolyPhen-2 0.21
- R46K (p.Arg46Lys), rs199920124, ClinGen CA196958120, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, CADD 21.20, PolyPhen-2 0.00, Uncertain significance, Hereditary fructosuria
- R46W (p.Arg46Trp), rs41281039, ClinGen CA129579, ClinVar RCV000023970, ClinVar RCV000728543, CADD 25.80, PolyPhen-2 0.89, Uncertain significance, ALDOB-related disorder; not specified; not provided
- I47S (p.Ile47Ser), Ensembl rs1831192961, CADD 28.40, PolyPhen-2 0.98
- K48N (p.Lys48Asn), TOPMed rs1420389591, CADD 15.90, PolyPhen-2 0.00, Uncertain significance, Hereditary fructosuria
- T52A (p.Thr52Ala), gnomAD rs1484672819, CADD 23.50, PolyPhen-2 0.34
- T52I (p.Thr52Ile), gnomAD rs1241120665, CADD 23.50, PolyPhen-2 0.40
- T52K (p.Thr52Lys), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- E53* (p.Glu53Ter), rs2490128994, ClinGen CA374265978, ClinVar RCV002309134, Likely pathogenic
- E54D (p.Glu54Asp), ExAC rs2854709, TOPMed rs2854709, gnomAD rs2854709, CADD 18.70, PolyPhen-2 0.11, Likely benign
- E54K (p.Glu54Lys), ExAC rs752642604, TOPMed rs752642604, gnomAD rs752642604, CADD 26.30, PolyPhen-2 0.72
- N55K (p.Asn55Lys), rs759273480, NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, ExAC rs759273480, CADD 23.50, PolyPhen-2 0.78, Likely benign
- N55T (p.Asn55Thr), Ensembl rs1588172355
- R56C (p.Arg56Cys), rs201397971, ClinGen CA5161711, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 32.00, PolyPhen-2 1.00, Uncertain significance, Inborn genetic diseases; Hereditary fructosuria
- R56H (p.Arg56His), rs200050226, ClinGen CA5161710, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 26.30, PolyPhen-2 1.00, Uncertain significance, Inborn genetic diseases
- R56L (p.Arg56Leu), rs200050226, ClinGen CA5161709, ClinVar RCV003258644, ExAC rs200050226, CADD 25.90, PolyPhen-2 0.93, Uncertain significance, Inborn genetic diseases
- R56P (p.Arg56Pro), ExAC rs200050226, TOPMed rs200050226, gnomAD rs200050226, CADD 27.40, PolyPhen-2 1.00, Uncertain significance
- R56S (p.Arg56Ser), ExAC rs201397971, TOPMed rs201397971, gnomAD rs201397971, CADD 28.20, PolyPhen-2 1.00, Uncertain significance
- R57L (p.Arg57Leu), rs370761101, ClinGen CA5161707, ClinVar RCV002712791, ESP rs370761101, AlphaMissense 0.99, MetaLR 0.87, Uncertain significance, Inborn genetic diseases
- R57P (p.Arg57Pro), rs370761101, ClinGen CA374265954, ClinVar RCV001376702, ESP rs370761101, AlphaMissense 0.99, MetaLR 0.87, Likely pathogenic, Hereditary fructosuria
- R57Q (p.Arg57Gln), ESP rs370761101, ExAC rs370761101, TOPMed rs370761101, gnomAD rs370761101, AlphaMissense 0.99, MetaLR 0.87, Likely pathogenic
- R57W (p.Arg57Trp), rs570143313, NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, 1000Genomes rs570143313, CADD 28.00, PolyPhen-2 1.00, Uncertain significance, ALDOB-related disorder
- Q58* (p.Gln58Ter), rs1831192129, ClinGen CA374265953, ClinVar RCV001263985, Ensembl rs1831192129, Likely pathogenic
- Q58R (p.Gln58Arg), TOPMed rs1831192095, CADD 19.80, PolyPhen-2 0.00
- F59L (p.Phe59Leu), ExAC rs777050401, gnomAD rs777050401, CADD 23.10, PolyPhen-2 0.07
- R60* (p.Arg60Ter), rs118204429, ClinGen CA339813, cosmic curated COSV66397, ClinVar RCV000000501, CADD 37.00, Pathogenic
- R60Q (p.Arg60Gln), rs141267935, ClinGen CA5161704, cosmic curated COSV66398, ClinVar RCV000731956, CADD 27.70, PolyPhen-2 0.95, Uncertain significance, Inborn genetic diseases; not provided; Hereditary fructosuria
- E61D (p.Glu61Asp), gnomAD rs1373617424, CADD 13.80, PolyPhen-2 0.02
- E61K (p.Glu61Lys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- I62L (p.Ile62Leu), Ensembl rs1588172330
- L63F (p.Leu63Phe), rs780352710, ClinGen CA5161703, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 26.60, PolyPhen-2 0.95, Uncertain significance, Hereditary fructosuria
- L63S (p.Leu63Ser), NCI-TCGA Cosmic COSV6639, Variant assessed as somatic; high impact.
- F64C (p.Phe64Cys), rs151219186, ESP rs151219186, TOPMed rs151219186, AlphaMissense 0.74, MetaLR 0.84, Variant assessed as somatic; moderate impact.
- F64L (p.Phe64Leu), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, Variant assessed as somatic; moderate impact.
- S65C (p.Ser65Cys), Ensembl rs1588172314
- S65F (p.Ser65Phe), NCI-TCGA Cosmic COSV1008, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, Variant assessed as somatic; moderate impact.
- S65T (p.Ser65Thr), Ensembl rs1588172318
- V66L (p.Val66Leu), ExAC rs772436722, TOPMed rs772436722, gnomAD rs772436722, CADD 17.70, PolyPhen-2 0.04
- V66M (p.Val66Met), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, CADD 22.50, PolyPhen-2 0.80, Variant assessed as somatic; moderate impact.
- S68C (p.Ser68Cys), ExAC rs746149471, gnomAD rs746149471, CADD 20.30, PolyPhen-2 0.01
- S68N (p.Ser68Asn), Ensembl rs1588172303
- I70F (p.Ile70Phe), ExAC rs757318986, TOPMed rs757318986, gnomAD rs757318986, CADD 8.72, PolyPhen-2 0.01
- I70T (p.Ile70Thr), rs752633158, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 26.90, PolyPhen-2 0.82, Variant assessed as somatic; moderate impact.
- N71K (p.Asn71Lys), TOPMed rs1831191065, gnomAD rs1831191065, CADD 19.70, PolyPhen-2 0.00, Uncertain significance, Inborn genetic diseases
- N71S (p.Asn71Ser), Ensembl rs1588172285, CADD 10.20, PolyPhen-2 0.00
- Q72* (p.Gln72Ter), rs1831191030, ClinGen CA374265861, ClinVar RCV001263984, Ensembl rs1831191030, Likely pathogenic
- S73I (p.Ser73Ile), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- I74T (p.Ile74Thr), rs781023784, ClinGen CA5161697, ClinVar RCV000666190, UniProt VAR 020822, CADD 25.60, PolyPhen-2 0.98, Conflicting interpretations, Hereditary fructosuria
- G75A (p.Gly75Ala), ESP rs375679562, ExAC rs375679562, TOPMed rs375679562, gnomAD rs375679562, CADD 22.60
- G75E (p.Gly75Glu), ESP rs375679562, ExAC rs375679562, TOPMed rs375679562, gnomAD rs375679562, CADD 23.00, PolyPhen-2 0.98, Uncertain significance, Inborn genetic diseases
- G75R (p.Gly75Arg), rs747604233, ClinGen CA5161695, cosmic curated COSV10971, ClinVar RCV002954646, CADD 24.40, PolyPhen-2 0.97, Uncertain significance, Hereditary fructosuria
- G76A (p.Gly76Ala), rs764779161, ClinGen CA5161691, ClinVar RCV004400683, ExAC rs764779161, CADD 23.90, PolyPhen-2 0.89, Uncertain significance, Inborn genetic diseases
- G76D (p.Gly76Asp), ExAC rs764779161, TOPMed rs764779161, gnomAD rs764779161, CADD 24.40, PolyPhen-2 0.98, Uncertain significance, Inborn genetic diseases
- G76S (p.Gly76Ser), rs759204107, ClinGen CA5161692, ClinVar RCV000592985, ClinVar RCV002532512, CADD 24.40, PolyPhen-2 1.00, Uncertain significance, Inborn genetic diseases; not provided; Hereditary fructosuria
- G76V (p.Gly76Val), rs764779161, ClinGen CA374265836, ClinVar RCV002248966, ExAC rs764779161, CADD 24.30, PolyPhen-2 1.00, Likely pathogenic, Hereditary fructosuria
- I78N (p.Ile78Asn), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, CADD 27.40, PolyPhen-2 1.00, Variant assessed as somatic; moderate impact.
- L79I (p.Leu79Ile), Ensembl rs1564078835, CADD 24.90, PolyPhen-2 0.92
- L79R (p.Leu79Arg), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, Variant assessed as somatic; moderate impact.
- H81Y (p.His81Tyr), Ensembl rs1831190571
- E82D (p.Glu82Asp), Ensembl rs1831190482
- E82K (p.Glu82Lys), cosmic curated COSV10442, ExAC rs777153196, TOPMed rs777153196, gnomAD rs777153196, CADD 27.60, PolyPhen-2 0.99, Uncertain significance, Inborn genetic diseases
- T83I (p.Thr83Ile), TOPMed rs568367333, gnomAD rs568367333, CADD 26.70, PolyPhen-2 1.00
- T83N (p.Thr83Asn), TOPMed rs568367333, gnomAD rs568367333, CADD 25.90, PolyPhen-2 1.00
- L84F (p.Leu84Phe), rs769043841, ClinGen CA5161688, ClinVar RCV003342557, ExAC rs769043841, CADD 22.60, PolyPhen-2 0.21, Uncertain significance, Inborn genetic diseases
- Y85* (p.Tyr85Ter), rs761063847, ClinGen CA374265776, ClinVar RCV002007182, ClinVar RCV002563614, Pathogenic
- Q86* (p.Gln86Ter), TOPMed rs1480911171
- Q86K (p.Gln86Lys), TOPMed rs1480911171, CADD 26.40
- Q86L (p.Gln86Leu), TOPMed rs1831190153, CADD 27.80, PolyPhen-2 0.99
- D88E (p.Asp88Glu), rs200585150, ClinGen CA5161686, ClinVar RCV000674895, ClinVar RCV000725650, CADD 20.80, PolyPhen-2 0.13, Conflicting interpretations, not specified; not provided; Hereditary fructosuria
- D88G (p.Asp88Gly), TOPMed rs1831190094, gnomAD rs1831190094, CADD 23.40, PolyPhen-2 0.04
- S89R (p.Ser89Arg), gnomAD rs1399264506
- Q90H (p.Gln90His), TOPMed rs1176960115, gnomAD rs1176960115, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, CADD 23.10, PolyPhen-2 0.00, Uncertain significance
- G91* (p.Gly91Ter), rs1831189846, ClinGen CA374265734, ClinVar RCV003597587, AlphaMissense 0.66, MetaLR 0.94, Pathogenic
- G91A (p.Gly91Ala), NCI-TCGA Cosmic COSV6639, Variant assessed as somatic; moderate impact.
- G91E (p.Gly91Glu), cosmic curated COSV66397, gnomAD rs1470738631, CADD 26.20, PolyPhen-2 0.95
- G91R (p.Gly91Arg), TOPMed rs1831189846, AlphaMissense 0.66, MetaLR 0.94
- K92M (p.Lys92Met), TOPMed rs1426817706, gnomAD rs1426817706, CADD 22.20, PolyPhen-2 0.14
- K92N (p.Lys92Asn), gnomAD rs1198275503, CADD 17.20, PolyPhen-2 0.35
- F94L (p.Phe94Leu), rs549682194, ClinGen CA5161685, ClinVar RCV004400689, ExAC rs549682194, CADD 21.70, PolyPhen-2 0.09, Uncertain significance, Inborn genetic diseases
- N96D (p.Asn96Asp), Ensembl rs1831189558
- N96I (p.Asn96Ile), TOPMed rs1479978704, gnomAD rs1479978704
- N96S (p.Asn96Ser), TOPMed rs1479978704, gnomAD rs1479978704, CADD 15.80, PolyPhen-2 0.00
- I97F (p.Ile97Phe), ExAC rs771004498, gnomAD rs771004498, CADD 18.80, PolyPhen-2 0.03
- I97N (p.Ile97Asn), gnomAD rs1204761318, CADD 27.40, PolyPhen-2 0.83
- I97T (p.Ile97Thr), gnomAD rs1204761318
- I97V (p.Ile97Val), ExAC rs771004498, gnomAD rs771004498, CADD 11.60, PolyPhen-2 0.00
- L98P (p.Leu98Pro), 1000Genomes rs200121991, gnomAD rs200121991
- K99E (p.Lys99Glu), rs781126536, ClinGen CA5161680, ClinVar RCV004400696, ExAC rs781126536, CADD 24.10, PolyPhen-2 0.21, Uncertain significance, Inborn genetic diseases
- K99N (p.Lys99Asn), ExAC rs754861661, gnomAD rs754861661, CADD 21.20, PolyPhen-2 0.23
- E100K (p.Glu100Lys), rs867022678, NCI-TCGA Cosmic COSV6639, cosmic curated COSV66397, Ensembl rs867022678, AlphaMissense 0.18, MetaLR 0.36, Variant assessed as somatic; moderate impact.
- K101N (p.Lys101Asn), TOPMed rs962536647, gnomAD rs962536647, CADD 18.00, PolyPhen-2 0.13
- G102E (p.Gly102Glu), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10087, Ensembl rs1831189050, Variant assessed as somatic; moderate impact.
- I103F (p.Ile103Phe), NCI-TCGA TCGA novel, CADD 31.00, PolyPhen-2 0.85, Variant assessed as somatic; moderate impact.
- V104L (p.Val104Leu), ExAC rs779797602, TOPMed rs779797602, gnomAD rs779797602
- V104M (p.Val104Met), cosmic curated COSV66398, ExAC rs779797602, TOPMed rs779797602, gnomAD rs779797602, CADD 24.10, PolyPhen-2 0.55
- V105G (p.Val105Gly), ExAC rs758242037, TOPMed rs758242037, gnomAD rs758242037, CADD 29.20, PolyPhen-2 0.98
- V105M (p.Val105Met), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, CADD 24.50, PolyPhen-2 0.82, Variant assessed as somatic; moderate impact.
- I107M (p.Ile107Met), gnomAD rs1403312459, CADD 24.50
- K108E (p.Lys108Glu), Ensembl rs1214506262
- L109* (p.Leu109Ter), gnomAD rs1264074747, CADD 41.00
- D110N (p.Asp110Asn), NCI-TCGA Cosmic COSV6639, cosmic curated COSV66398, Variant assessed as somatic; moderate impact.
- D110V (p.Asp110Val), gnomAD rs1203633267, CADD 27.60, PolyPhen-2 0.87
- Q111* (p.Gln111Ter), rs528914024, ClinGen CA196957692, ClinVar RCV001376703, 1000Genomes rs528914024, CADD 41.00, Pathogenic
- Q111R (p.Gln111Arg), gnomAD rs1210158463, CADD 23.90, PolyPhen-2 0.00
- G112R (p.Gly112Arg), rs373330514, ClinGen CA5161651, ClinVar RCV000729970, ClinVar RCV002533115, CADD 28.90, PolyPhen-2 0.98, Uncertain significance, not provided; Inborn genetic diseases; Hereditary fructosuria
- G113D (p.Gly113Asp), Ensembl rs2118358776, CADD 6.22, PolyPhen-2 0.00
Public ALDOB analysis runs
- ALDOB analysis run — ALDOB (814 variants) — completed 2026-08-21