TGM1 (P22735) variants and mutations
TGM1 (also known as P22735) is a human protein-coding gene encoding a protein-glutamine gamma-glutamyltransferase K protein. It crosslinks structural proteins and lipids during formation of the cornified envelope, creating the mechanically resilient outer skin barrier. Biallelic loss-of-function variants are a major cause of autosomal recessive congenital ichthyosis, particularly lamellar ichthyosis. This analysis covers 1,372 TGM1 variants and mutations. Of these, 78% have computational variant effect predictions. Disease context includes lamellar ichthyosis, autosomal recessive congenital ichthyosis, and congenital reticular ichthyosiform erythroderma. Example TGM1 variants include M1?, M1V, and D3G.
Variant analysis overview
- Gene: TGM1
- Protein: P22735
- UniProt accession: P22735
- Organism: Homo sapiens
- Variants analyzed: 1372
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 1,104 unspecified-consequence records; 122 missense variants; 13 frameshift variants; 112 synonymous variants; 2 in-frame deletions; 7 stop-gained variants; 1 stop lost; 3 splice-region variants; 1 in-frame insertions; 8 substitution
- Prediction scores: 1,077 variants have prediction scores (78% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: lamellar ichthyosis, autosomal recessive congenital ichthyosis, congenital reticular ichthyosiform erythroderma, Abnormality of the skin, ichthyosis, congenital non-bullous ichthyosiform erythroderma, acral self-healing collodion baby, bathing suit ichthyosis, self-healing collodion baby, inherited ichthyosis, Treacher Collins syndrome 1, neurodegenerative disease.
Protein structure and variant hotspots
- Protein features: 10 binding sites; 7 post-translational modification sites.
- PTM context: 14 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable TGM1 variants
Examples include M1?, M1V, D3G, P5L, P5S, R6C, R6H, R6L. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1?, NCI-TCGA Cosmic COSV5286, Variant assessed as somatic; high impact.
- M1V (p.Met1Val), rs760172387, ClinGen CA7131570, ClinVar RCV001110690, MetaLR 0.32, MetaSVM -0.82, Uncertain significance, Autosomal recessive congenital ichthyosis 1
- D3G (p.Asp3Gly), TOPMed rs1441749745, gnomAD rs1441749745, REVEL 0.37, CADD 24.40
- P5L (p.Pro5Leu), Ensembl rs2040821450
- P5S (p.Pro5Ser), gnomAD rs1289089282, REVEL 0.41, CADD 15.00
- R6C (p.Arg6Cys), rs372412279, ESP rs372412279, TOPMed rs372412279, gnomAD rs372412279, REVEL 0.45, CADD 24.20, Uncertain significance, Autosomal recessive congenital ichthyosis 1; Inborn genetic diseases
- R6H (p.Arg6His), rs368781510, ESP rs368781510, TOPMed rs368781510, gnomAD rs368781510, REVEL 0.43, CADD 24.00, Variant assessed as somatic; moderate impact.
- R6L (p.Arg6Leu), ESP rs368781510, TOPMed rs368781510, gnomAD rs368781510
- S7P (p.Ser7Pro), Ensembl rs2139028795
- D8H (p.Asp8His), 1000Genomes rs376706308, ESP rs376706308, ExAC rs376706308, TOPMed rs376706308, REVEL 0.39, CADD 23.90, Uncertain significance, Inborn genetic diseases
- D8N (p.Asp8Asn), 1000Genomes rs376706308, ESP rs376706308, ExAC rs376706308, TOPMed rs376706308, REVEL 0.28, CADD 23.50
- V9G (p.Val9Gly), ExAC rs267603965, gnomAD rs267603965, REVEL 0.44, CADD 18.50
- V9M (p.Val9Met), Ensembl rs2040821278, NCI-TCGA Cosmic COSV9925, Variant assessed as somatic; moderate impact.
- G10V (p.Gly10Val), gnomAD rs2040821232, REVEL 0.48, CADD 23.40
- R11C (p.Arg11Cys), ExAC rs747931513, TOPMed rs747931513, gnomAD rs747931513, REVEL 0.48, CADD 25.70
- R11H (p.Arg11His), rs764819314, ExAC rs764819314, TOPMed rs764819314, gnomAD rs764819314, REVEL 0.43, CADD 24.30, Uncertain significance, Inborn genetic diseases
- R11S (p.Arg11Ser), ExAC rs747931513, TOPMed rs747931513, gnomAD rs747931513, REVEL 0.43, CADD 24.50
- W12* (p.Trp12Ter), rs2040821117, gnomAD rs2040821117, ClinGen CA389282857, ClinVar RCV003064190, CADD 36.00, Pathogenic
- W12C (p.Trp12Cys), TOPMed rs2040821099
- W12R (p.Trp12Arg), gnomAD rs1413293925, REVEL 0.45, CADD 24.40, Uncertain significance, Inborn genetic diseases
- G13D (p.Gly13Asp), gnomAD rs1164800116, REVEL 0.40, CADD 17.40
- G13S (p.Gly13Ser), TOPMed rs2040821081
- G14D (p.Gly14Asp), gnomAD rs1473968359, REVEL 0.43, CADD 14.40
- G14S (p.Gly14Ser), TOPMed rs2040821007
- P16R (p.Pro16Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L17V (p.Leu17Val), gnomAD rs1258993099, REVEL 0.37, CADD 9.55
- P19H (p.Pro19His), TOPMed rs1321365902, gnomAD rs1321365902, REVEL 0.37, CADD 23.10
- P19L (p.Pro19Leu), TOPMed rs1321365902, gnomAD rs1321365902, REVEL 0.39, CADD 23.30
- P19T (p.Pro19Thr), TOPMed rs919743006
- P20A (p.Pro20Ala), TOPMed rs1297093834, gnomAD rs1297093834, REVEL 0.38, CADD 4.80
- P20L (p.Pro20Leu), rs1445996067, gnomAD rs1445996067, AlphaMissense 0.09, MetaLR 0.32, Variant assessed as somatic; moderate impact.
- P20S (p.Pro20Ser), TOPMed rs1297093834, gnomAD rs1297093834, REVEL 0.35, CADD 7.15
- T21A (p.Thr21Ala), rs140542428, 1000Genomes rs140542428, ESP rs140542428, ExAC rs140542428, REVEL 0.26, CADD 0.55, Conflicting interpretations, not provided; Inborn genetic diseases; Autosomal recessive congenital ichthyosis
- T21I (p.Thr21Ile), TOPMed rs2040820632, Uncertain significance, Inborn genetic diseases
- T21S (p.Thr21Ser), 1000Genomes rs140542428, ESP rs140542428, ExAC rs140542428, TOPMed rs140542428, REVEL 0.23, CADD 1.62, Likely benign
- T22A (p.Thr22Ala), gnomAD rs1272511953
- T22M (p.Thr22Met), rs201774398, ESP rs201774398, ExAC rs201774398, TOPMed rs201774398, REVEL 0.33, CADD 22.40, Conflicting interpretations, Inborn genetic diseases; not provided
- T22R (p.Thr22Arg), ESP rs201774398, ExAC rs201774398, TOPMed rs201774398, gnomAD rs201774398, Likely benign
- P23A (p.Pro23Ala), TOPMed rs1286022002, gnomAD rs1286022002, REVEL 0.27, CADD 16.70
- P23Q (p.Pro23Gln), TOPMed rs1019810397, gnomAD rs1019810397, REVEL 0.35, CADD 22.50, Uncertain significance, Autosomal recessive congenital ichthyosis 1
- S24C (p.Ser24Cys), NCI-TCGA Cosmic COSV5286, Variant assessed as somatic; moderate impact.
- S24F (p.Ser24Phe), gnomAD rs1245797682, REVEL 0.35, CADD 24.60, Uncertain significance, Inborn genetic diseases
- P25L (p.Pro25Leu), TOPMed rs1463129797, gnomAD rs1463129797, REVEL 0.32, CADD 22.20
- P25S (p.Pro25Ser), ExAC rs753092145, gnomAD rs753092145, REVEL 0.33, CADD 20.40
- E26G (p.Glu26Gly), TOPMed rs2040820316, gnomAD rs2040820316, REVEL 0.34, CADD 23.20, Uncertain significance, Autosomal recessive congenital ichthyosis 1
- P27L (p.Pro27Leu), Ensembl rs1008918554, REVEL 0.37, CADD 22.90
- P27S (p.Pro27Ser), gnomAD rs1384319244
- E28* (p.Glu28Ter), ExAC rs760012789, TOPMed rs760012789, gnomAD rs760012789, CADD 36.00
- E28A (p.Glu28Ala), gnomAD rs1325894326, REVEL 0.27, CADD 22.20
- E28D (p.Glu28Asp), gnomAD rs1460335965, REVEL 0.44, CADD 9.44
- E28K (p.Glu28Lys), ExAC rs760012789, TOPMed rs760012789, gnomAD rs760012789, REVEL 0.41, CADD 21.10
- E28Q (p.Glu28Gln), ExAC rs760012789, TOPMed rs760012789, gnomAD rs760012789, REVEL 0.35, CADD 14.30
- P29A (p.Pro29Ala), gnomAD rs1419399482, REVEL 0.26, CADD 18.90
- P29L (p.Pro29Leu), TOPMed rs200873762, gnomAD rs200873762, REVEL 0.30, CADD 22.40
- D32E (p.Asp32Glu), 1000Genomes rs151333205, ESP rs151333205, TOPMed rs151333205, gnomAD rs151333205, REVEL 0.26, CADD 7.04, Likely benign
- D32H (p.Asp32His), TOPMed rs1474889585, gnomAD rs1474889585
- D32N (p.Asp32Asn), TOPMed rs1474889585, gnomAD rs1474889585, REVEL 0.28, CADD 15.50
- G33E (p.Gly33Glu), Ensembl rs2139028595
- G33R (p.Gly33Arg), rs142455594, ESP rs142455594, ExAC rs142455594, TOPMed rs142455594, REVEL 0.29, CADD 6.17, Conflicting interpretations, not provided; Autosomal recessive congenital ichthyosis 1; Inborn genetic diseas
- R34C (p.Arg34Cys), rs149148326, ClinGen CA7131546, ClinVar RCV001277605, ClinVar RCV002537754, REVEL 0.39, CADD 22.90, Conflicting interpretations, not provided; Autosomal recessive congenital ichthyosis 1
- R34H (p.Arg34His), TOPMed rs1449897250, gnomAD rs1449897250, REVEL 0.28, CADD 12.90
- R34P (p.Arg34Pro), TOPMed rs1449897250, gnomAD rs1449897250, REVEL 0.40, CADD 17.90
- S35C (p.Ser35Cys), TOPMed rs1211811598, gnomAD rs1211811598, REVEL 0.28, CADD 12.30
- S35F (p.Ser35Phe), TOPMed rs1211811598, gnomAD rs1211811598, REVEL 0.31, CADD 12.30
- R36C (p.Arg36Cys), 1000Genomes rs145197904, ESP rs145197904, ExAC rs145197904, TOPMed rs145197904, REVEL 0.49, CADD 19.10, Uncertain significance, Inborn genetic diseases
- R36G (p.Arg36Gly), 1000Genomes rs145197904, ESP rs145197904, ExAC rs145197904, TOPMed rs145197904, REVEL 0.46, CADD 12.10, Likely benign
- R36H (p.Arg36His), rs367872941, ClinGen CA7131543, ClinVar RCV002616844, ClinVar RCV005505604, REVEL 0.34, CADD 17.20, Conflicting interpretations, Inborn genetic diseases; not provided
- R36L (p.Arg36Leu), ESP rs367872941, ExAC rs367872941, TOPMed rs367872941, gnomAD rs367872941, REVEL 0.47, CADD 16.90, Likely benign
- R36S (p.Arg36Ser), rs145197904, ClinGen CA7131544, ClinVar RCV000896031, ClinVar RCV001110686, REVEL 0.47, CADD 10.00, Conflicting interpretations, Inborn genetic diseases; not provided; not specified
- R37K (p.Arg37Lys), TOPMed rs1344562454, gnomAD rs1344562454, REVEL 0.15, CADD 10.30
- G38* (p.Gly38Ter), TOPMed rs1268694454, gnomAD rs1268694454
- G38R (p.Gly38Arg), TOPMed rs1268694454, gnomAD rs1268694454, REVEL 0.28, CADD 16.10
- G40S (p.Gly40Ser), Ensembl rs2040819651, REVEL 0.21, CADD 8.45
- R41C (p.Arg41Cys), rs776286185, NCI-TCGA Cosmic COSV5286, ExAC rs776286185, TOPMed rs776286185, REVEL 0.47, CADD 23.00, Variant assessed as somatic; moderate impact.
- R41H (p.Arg41His), rs768398275, ExAC rs768398275, TOPMed rs768398275, gnomAD rs768398275, REVEL 0.39, CADD 24.50, Uncertain significance, Inborn genetic diseases; Autosomal recessive congenital ichthyosis 1
- S42A (p.Ser42Ala), Ensembl rs1566381476, REVEL 0.30, CADD 13.50
- S42C (p.Ser42Cys), 1000Genomes rs41295338, ESP rs41295338, ExAC rs41295338, TOPMed rs41295338, REVEL 0.50, CADD 24.00, Benign, in ARCI1
- S42Y (p.Ser42Tyr), rs41295338, 1000Genomes rs41295338, ESP rs41295338, ExAC rs41295338, REVEL 0.56, CADD 23.80, Conflicting interpretations, not specified; not provided; Autosomal recessive congenital ichthyosis 1
- W44* (p.Trp44Ter), rs886039654, ClinGen CA10588573, ClinVar RCV000255767, ClinVar RCV000666492, CADD 37.00, Pathogenic
- W44R (p.Trp44Arg), TOPMed rs887095058, gnomAD rs887095058, REVEL 0.58, CADD 25.80
- W44fsX, rs886039654, Likely pathogenic / Pathogenic
- A45S (p.Ala45Ser), TOPMed rs1444351615, gnomAD rs1444351615, REVEL 0.32, CADD 20.10
- R46C (p.Arg46Cys), rs752411526, ClinGen CA7131537, ClinVar RCV004474564, ExAC rs752411526, REVEL 0.67, CADD 26.10, Uncertain significance, Inborn genetic diseases
- R46H (p.Arg46His), rs777960926, ExAC rs777960926, TOPMed rs777960926, gnomAD rs777960926, REVEL 0.55, CADD 24.20, Variant assessed as somatic; moderate impact.
- R46L (p.Arg46Leu), ExAC rs777960926, TOPMed rs777960926, gnomAD rs777960926, REVEL 0.61, CADD 25.80, Uncertain significance, Inborn genetic diseases
- C48Y (p.Cys48Tyr), ExAC rs756287272, gnomAD rs756287272, REVEL 0.54, CADD 23.70
- G49D (p.Gly49Asp), rs1169342293, TOPMed rs1169342293, gnomAD rs1169342293, REVEL 0.34, CADD 14.90, Uncertain significance, Inborn genetic diseases
- C50W (p.Cys50Trp), ExAC rs781571049, gnomAD rs781571049, REVEL 0.57, CADD 25.10
- C50Y (p.Cys50Tyr), TOPMed rs2040819294, gnomAD rs2040819294, REVEL 0.64, CADD 24.80, Uncertain significance, Autosomal recessive congenital ichthyosis 1
- C51R (p.Cys51Arg), TOPMed rs1566381437, gnomAD rs1566381437, REVEL 0.72, CADD 25.00
- C51S (p.Cys51Ser), TOPMed rs1566381437, gnomAD rs1566381437, REVEL 0.71, CADD 24.50
- C53* (p.Cys53Ter), rs201432046, ClinGen CA257902252, ClinVar RCV000672592, TOPMed rs201432046, Likely pathogenic, in ARCI1
- C53S (p.Cys53Ser), UniProt VAR 058638, Pathogenic, in ARCI1
- R54* (p.Arg54Ter), rs140000324, 1000Genomes rs140000324, ESP rs140000324, ExAC rs140000324, CADD 34.00, Pathogenic
- R54G (p.Arg54Gly), 1000Genomes rs140000324, ESP rs140000324, ExAC rs140000324, TOPMed rs140000324, REVEL 0.29, CADD 15.00, Pathogenic
- R54L (p.Arg54Leu), 1000Genomes rs536915231, ExAC rs536915231, TOPMed rs536915231, gnomAD rs536915231, REVEL 0.41, CADD 19.00, Uncertain significance, Inborn genetic diseases
- R54Q (p.Arg54Gln), rs536915231, 1000Genomes rs536915231, ExAC rs536915231, TOPMed rs536915231, REVEL 0.19, CADD 14.90, Uncertain significance, Inborn genetic diseases
- A56E (p.Ala56Glu), 1000Genomes rs147479810, ESP rs147479810, ExAC rs147479810, TOPMed rs147479810, REVEL 0.38, CADD 0.02, Likely benign
- A56V (p.Ala56Val), rs147479810, ClinGen CA7131528, ClinVar RCV000907290, ClinVar RCV001109899, REVEL 0.33, CADD 0.20, Conflicting interpretations, Autosomal recessive congenital ichthyosis 1; not provided
- A57T (p.Ala57Thr), Ensembl rs867320439
- A57V (p.Ala57Val), gnomAD rs1437379232, REVEL 0.37, CADD 1.04, Uncertain significance, Inborn genetic diseases
- D58H (p.Asp58His), ESP rs139569235, ExAC rs139569235, TOPMed rs139569235, gnomAD rs139569235, REVEL 0.40, CADD 23.20
- D58Y (p.Asp58Tyr), ESP rs139569235, ExAC rs139569235, TOPMed rs139569235, gnomAD rs139569235, REVEL 0.42, CADD 23.30
- D60E (p.Asp60Glu), ExAC rs760445319, TOPMed rs760445319, gnomAD rs760445319, REVEL 0.30, CADD 24.00
- D60N (p.Asp60Asn), ExAC rs768306663, TOPMed rs768306663, gnomAD rs768306663, REVEL 0.30, CADD 23.60
- W61* (p.Trp61Ter), rs1232497911, gnomAD rs1232497911, ClinGen CA389280799, ClinVar RCV002908939, CADD 36.00, Pathogenic
- W61C (p.Trp61Cys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G62* (p.Gly62Ter), rs886041950, gnomAD rs886041950, ClinGen CA10603315, ClinVar RCV000285634, CADD 37.00, Pathogenic
- G62A (p.Gly62Ala), TOPMed rs2040818800, gnomAD rs2040818800
- G62E (p.Gly62Glu), TOPMed rs2040818800, gnomAD rs2040818800, REVEL 0.34, CADD 22.20
- P63H (p.Pro63His), ExAC rs775398833, gnomAD rs775398833, REVEL 0.26, CADD 15.60
- E64K (p.Glu64Lys), TOPMed rs2040818703
- P65H (p.Pro65His), TOPMed rs2040818663
- P65T (p.Pro65Thr), TOPMed rs1291960319
- S66T (p.Ser66Thr), gnomAD rs1442094581
- D67A (p.Asp67Ala), TOPMed rs1410259199
- S68A (p.Ser68Ala), rs778749307, ExAC rs778749307, TOPMed rs778749307, gnomAD rs778749307, REVEL 0.26, CADD 15.30, Uncertain significance, Inborn genetic diseases
- S68T (p.Ser68Thr), ExAC rs778749307, TOPMed rs778749307, gnomAD rs778749307, REVEL 0.25, CADD 15.20, Uncertain significance
- R69G (p.Arg69Gly), ExAC rs769930720, gnomAD rs769930720, REVEL 0.33, CADD 20.10, Uncertain significance, Inborn genetic diseases
- G70D (p.Gly70Asp), ExAC rs781552476, TOPMed rs781552476, gnomAD rs781552476, REVEL 0.20, CADD 1.04
- G70R (p.Gly70Arg), ESP rs150599652, ExAC rs150599652, TOPMed rs150599652, gnomAD rs150599652, REVEL 0.14, CADD 10.00, Uncertain significance, Autosomal recessive congenital ichthyosis 1
- G70S (p.Gly70Ser), rs150599652, ESP rs150599652, ExAC rs150599652, TOPMed rs150599652, REVEL 0.10, CADD 6.55, Conflicting interpretations, Inborn genetic diseases; not provided
- G70V (p.Gly70Val), ExAC rs781552476, TOPMed rs781552476, gnomAD rs781552476, NCI-TCGA TCGA novel, REVEL 0.12, CADD 3.46, Variant assessed as somatic; high impact.
- R71* (p.Arg71Ter), rs2040818118, Ensembl rs2040818118, ClinGen CA389280369, ClinVar RCV001387569, CADD 36.00, Pathogenic
- R71L (p.Arg71Leu), ESP rs374035643, ExAC rs374035643, TOPMed rs374035643, gnomAD rs374035643
- R71Q (p.Arg71Gln), ESP rs374035643, ExAC rs374035643, TOPMed rs374035643, gnomAD rs374035643, REVEL 0.23, CADD 16.60, Uncertain significance, Inborn genetic diseases
- S74I (p.Ser74Ile), ExAC rs750901013, gnomAD rs750901013
- S74R (p.Ser74Arg), 1000Genomes rs565811853, ExAC rs565811853, TOPMed rs565811853, gnomAD rs565811853, REVEL 0.23, CADD 5.85, Uncertain significance, Inborn genetic diseases
- S75A (p.Ser75Ala), ExAC rs761252462, gnomAD rs761252462, REVEL 0.27, CADD 1.82
- S75C (p.Ser75Cys), ExAC rs753400612, gnomAD rs753400612
- S75F (p.Ser75Phe), ExAC rs753400612, gnomAD rs753400612
- S75Y (p.Ser75Tyr), NCI-TCGA Cosmic COSV5286, Variant assessed as somatic; moderate impact.
- G76D (p.Gly76Asp), TOPMed rs1279774123, gnomAD rs1279774123
- G76S (p.Gly76Ser), ESP rs372349270, ExAC rs372349270, TOPMed rs372349270, gnomAD rs372349270, REVEL 0.16, CADD 7.33
- T77I (p.Thr77Ile), TOPMed rs1413403334, gnomAD rs1413403334, REVEL 0.18, CADD 1.29
- R78* (p.Arg78Ter), rs760429286, ExAC rs760429286, TOPMed rs760429286, gnomAD rs760429286, CADD 35.00, Pathogenic
- R78Q (p.Arg78Gln), rs775030916, ExAC rs775030916, TOPMed rs775030916, gnomAD rs775030916, REVEL 0.19, CADD 16.70, Variant assessed as somatic; moderate impact.
- R79I (p.Arg79Ile), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R79S (p.Arg79Ser), Ensembl rs1594574474
- P80H (p.Pro80His), ExAC rs767307328, TOPMed rs767307328, gnomAD rs767307328
- P80L (p.Pro80Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P80R (p.Pro80Arg), ExAC rs767307328, TOPMed rs767307328, gnomAD rs767307328, REVEL 0.23, CADD 20.80, Uncertain significance, Inborn genetic diseases
- P80S (p.Pro80Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G81V (p.Gly81Val), gnomAD rs1354248672, REVEL 0.20, CADD 0.43
- S82F (p.Ser82Phe), rs141792428, 1000Genomes rs141792428, ESP rs141792428, ExAC rs141792428, REVEL 0.32, CADD 23.20, Likely benign, not provided
- R83Q (p.Arg83Gln), rs771051927, ExAC rs771051927, TOPMed rs771051927, gnomAD rs771051927, REVEL 0.32, CADD 19.30, Conflicting interpretations, Inborn genetic diseases; not provided; not specified
- R83W (p.Arg83Trp), rs774288859, ClinGen CA7131501, ClinVar RCV003073708, ClinVar RCV004070224, REVEL 0.38, CADD 23.30, Conflicting interpretations, not provided; Inborn genetic diseases
- G84A (p.Gly84Ala), ExAC rs748234923, TOPMed rs748234923, gnomAD rs748234923, REVEL 0.16, CADD 12.30, Uncertain significance
- G84C (p.Gly84Cys), TOPMed rs1430637159, gnomAD rs1430637159, REVEL 0.24, CADD 21.70
- G84D (p.Gly84Asp), ExAC rs748234923, TOPMed rs748234923, gnomAD rs748234923, Uncertain significance, Inborn genetic diseases
- G84R (p.Gly84Arg), TOPMed rs1430637159, gnomAD rs1430637159
- G84V (p.Gly84Val), ExAC rs748234923, TOPMed rs748234923, gnomAD rs748234923, REVEL 0.13, CADD 14.70, Uncertain significance
- S85* (p.Ser85Ter), rs1441391864, ClinGen CA389279946, ClinVar RCV003474092, AlphaMissense 0.10, MetaLR 0.29, Likely pathogenic
- S85L (p.Ser85Leu), TOPMed rs1441391864, REVEL 0.14, AlphaMissense 0.10
- S85T (p.Ser85Thr), TOPMed rs987272366, gnomAD rs987272366, REVEL 0.16, CADD 7.51
- D86A (p.Asp86Ala), Ensembl rs1594574435
- S87F (p.Ser87Phe), Ensembl rs2040817394, REVEL 0.23, CADD 13.50
- S87P (p.Ser87Pro), Ensembl rs1594574395
- R88C (p.Arg88Cys), ExAC rs768743174, TOPMed rs768743174, gnomAD rs768743174, REVEL 0.28, CADD 20.40
- R88H (p.Arg88His), TOPMed rs1056539762, gnomAD rs1056539762, REVEL 0.11, CADD 8.95
- R88L (p.Arg88Leu), TOPMed rs1056539762, gnomAD rs1056539762
- R89Q (p.Arg89Gln), rs141492969, ClinGen CA7131495, ClinVar RCV001277602, ESP rs141492969, REVEL 0.22, CADD 1.11, Uncertain significance, Autosomal recessive congenital ichthyosis 1
- R89W (p.Arg89Trp), rs146189995, ClinGen CA7131496, ClinVar RCV001109897, ClinVar RCV004032147, REVEL 0.44, CADD 16.50, Uncertain significance, Inborn genetic diseases; not provided; Autosomal recessive congenital ichthyosis
- P90A (p.Pro90Ala), TOPMed rs1277230238, gnomAD rs1277230238, REVEL 0.28, CADD 16.90
- V91A (p.Val91Ala), rs1484506489, TOPMed rs1484506489, gnomAD rs1484506489, REVEL 0.18, CADD 0.09, Variant assessed as somatic; moderate impact.
- V91G (p.Val91Gly), TOPMed rs1484506489, gnomAD rs1484506489
- V91L (p.Val91Leu), rs779376697, ClinGen CA7131492, ClinVar RCV003274575, ExAC rs779376697, REVEL 0.13, CADD 0.61, Uncertain significance, Inborn genetic diseases
- S92A (p.Ser92Ala), gnomAD rs1270631760, REVEL 0.32, CADD 18.60
- S92F (p.Ser92Phe), NCI-TCGA Cosmic COSV5286, Variant assessed as somatic; moderate impact.
- S92T (p.Ser92Thr), gnomAD rs1270631760, REVEL 0.40, CADD 16.30
- R93Q (p.Arg93Gln), rs753328770, ExAC rs753328770, TOPMed rs753328770, gnomAD rs753328770, REVEL 0.35, CADD 21.20, Uncertain significance, Autosomal recessive congenital ichthyosis 1
- R93W (p.Arg93Trp), ExAC rs757823355, TOPMed rs757823355, gnomAD rs757823355, REVEL 0.47, CADD 22.80
- G94D (p.Gly94Asp), rs121918729, 1000Genomes rs121918729, ExAC rs121918729, TOPMed rs121918729, REVEL 0.58, CADD 13.40, Conflicting interpretations, not provided; Autosomal recessive congenital ichthyosis 1
- G96R (p.Gly96Arg), 1000Genomes rs547714904, ExAC rs547714904, TOPMed rs547714904, gnomAD rs547714904, REVEL 0.46, CADD 8.53
- G96S (p.Gly96Ser), rs547714904, 1000Genomes rs547714904, ExAC rs547714904, TOPMed rs547714904, REVEL 0.25, CADD 6.76, Variant assessed as somatic; moderate impact.
- V97A (p.Val97Ala), NCI-TCGA TCGA novel, TOPMed rs2040816323, Variant assessed as somatic; moderate impact.
- N98S (p.Asn98Ser), TOPMed rs575342998, gnomAD rs575342998, REVEL 0.24, CADD 13.80
- A99T (p.Ala99Thr), Ensembl rs2040816245
- G101R (p.Gly101Arg), TOPMed rs1321204183, gnomAD rs1321204183, REVEL 0.44, CADD 19.90
- G101V (p.Gly101Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
Public TGM1 analysis runs
- TGM1 analysis run — TGM1 (1,372 variants) — completed 2026-08-21