SPAST (Spastin) variants and mutations
SPAST (also known as Spastin) is a human protein-coding gene encoding a spastin protein. It severs microtubules and remodels the axonal cytoskeleton, enabling organelle transport and maintenance of very long corticospinal axons. Dominant loss-of-function variants are the most common cause of hereditary spastic paraplegia, classically SPG4. This analysis covers 1,384 SPAST variants and mutations. Of these, 80% have computational variant effect predictions. Disease context includes Autosomal dominant spastic paraplegia type 4, hereditary spastic paraplegia 4, and hereditary spastic paraplegia. Example SPAST variants include M1I, M1V, and N2S.
Variant analysis overview
- Gene: SPAST
- Protein: Spastin
- UniProt accession: Q9UBP0
- Organism: Homo sapiens
- Variants analyzed: 1384
- Variant scope: all variants
- Completed: 2026-08-22
Variant and mutation evidence
- Variant composition: 1,068 unspecified-consequence records; 115 synonymous variants; 173 missense variants; 8 frameshift variants; 4 stop-gained variants; 10 in-frame deletions; 1 in-frame insertions; 1 splice-region variants; 8 substitution
- Prediction scores: 1,110 variants have prediction scores (80% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Autosomal dominant spastic paraplegia type 4, hereditary spastic paraplegia 4, hereditary spastic paraplegia, Spastic paraplegia, Rare hereditary ataxia, hereditary disease, hereditary ataxia, Spastic paraparesis, Tip-toe gait, Spasticity, neurodevelopmental disorder, cerebral palsy.
Protein structure and variant hotspots
- Protein features: 1 domains; 1 binding sites; 4 post-translational modification sites.
- Structural context: 186 variants have structural context.
- PTM context: 7 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable SPAST variants
Examples include M1I, M1V, N2S, S3F, S3Y, S3S, P4A, P4L. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1I (p.Met1Ile), rs1676383079, ClinGen CA346601174, ClinVar RCV002598340, MetaLR 0.74, MetaSVM 0.46, Uncertain significance, Hereditary spastic paraplegia 4
- M1V (p.Met1Val), rs2465679256, ClinGen CA346601167, ClinVar RCV003415541, ClinVar RCV003484419, Uncertain significance, Hereditary spastic paraplegia 4; not provided
- N2S (p.Asn2Ser), gnomAD rs1230051542, REVEL 0.19, CADD 18.40
- S3F (p.Ser3Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S3Y (p.Ser3Tyr), gnomAD rs1271058224, REVEL 0.46, CADD 26.60
- S3S (p.Ser3Ser), gnomAD 2-32063840-T-C, CADD 15.50
- P4A (p.Pro4Ala), rs937319046, ClinGen CA346601190, ClinVar RCV001848141, TOPMed rs937319046, REVEL 0.43, CADD 23.20, Uncertain significance, Hereditary spastic paraplegia
- P4L (p.Pro4Leu), ExAC rs751225341, gnomAD rs751225341, REVEL 0.44, CADD 24.00, Uncertain significance
- P4R (p.Pro4Arg), rs751225341, ClinGen CA1600449, ClinVar RCV002933161, ClinVar RCV004774760, REVEL 0.54, CADD 25.90, Uncertain significance, not provided; Hereditary spastic paraplegia 4
- P4S (p.Pro4Ser), rs937319046, ClinGen CA45201382, ClinVar RCV002261678, ClinVar RCV003774805, REVEL 0.47, CADD 23.70, Uncertain significance, Hereditary spastic paraplegia 4; not provided
- P4T (p.Pro4Thr), gnomAD 2-32063841-C-A, REVEL 0.45, CADD 23.50
- P4Q (p.Pro4Gln), gnomAD 2-32063842-C-A, REVEL 0.51, CADD 25.80
- P4P (p.Pro4Pro), rs759236371, gnomAD 2-32063843-G-T, CADD 14.10
- G5D (p.Gly5Asp), TOPMed rs1356764866, REVEL 0.42, CADD 22.80
- G5V (p.Gly5Val), gnomAD 2-32063842-CG-C, CADD 24.90
- G5R (p.Gly5Arg), gnomAD 2-32063844-G-C, REVEL 0.38, CADD 24.70
- G5S (p.Gly5Ser), gnomAD 2-32063844-G-A, REVEL 0.34, CADD 24.30
- G5C (p.Gly5Cys), gnomAD 2-32063844-G-T, REVEL 0.42, CADD 25.20
- G5G (p.Gly5Gly), rs754256093, gnomAD 2-32063846-T-G, CADD 13.90
- G6* (p.Gly6Ter), rs2465679369, ClinGen CA346601200, ClinVar RCV003633041, CADD 37.00, Pathogenic
- G6E (p.Gly6Glu), rs757518655, ClinGen CA1600453, ClinVar RCV003063839, ExAC rs757518655, REVEL 0.41, CADD 24.20, Uncertain significance, Hereditary spastic paraplegia 4
- G6D (p.Gly6Asp), gnomAD 2-32063846-TG-T, CADD 29.10
- G6V (p.Gly6Val), gnomAD 2-32063848-G-T, REVEL 0.44, CADD 24.40
- G6G (p.Gly6Gly), gnomAD 2-32063849-A-G, CADD 16.20
- R7L (p.Arg7Leu), rs750900931, ClinGen CA1600455, ClinVar RCV001931590, ExAC rs750900931, REVEL 0.55, CADD 25.20, Uncertain significance, Hereditary spastic paraplegia 4
- R7P (p.Arg7Pro), rs750900931, ClinGen CA1600456, ClinVar RCV001897865, ExAC rs750900931, REVEL 0.56, CADD 25.80, Uncertain significance, Hereditary spastic paraplegia 4
- R7Q (p.Arg7Gln), NCI-TCGA TCGA novel, REVEL 0.40, CADD 25.10, Variant assessed as somatic; moderate impact.
- R7* (p.Arg7Ter), gnomAD 2-32063850-C-T, CADD 36.00
- R7R (p.Arg7Arg), rs779449573, gnomAD 2-32063850-C-A, CADD 15.10
- G8E (p.Gly8Glu), rs1477506013, ClinGen CA346601209, ClinVar RCV003860963, TOPMed rs1477506013, REVEL 0.30, CADD 22.90, Uncertain significance, Hereditary spastic paraplegia 4
- G8R (p.Gly8Arg), TOPMed rs950926374, gnomAD rs950926374, REVEL 0.30, CADD 20.80
- G8W (p.Gly8Trp), gnomAD 2-32063853-G-T, REVEL 0.31, CADD 23.50
- G8G (p.Gly8Gly), gnomAD 2-32063855-G-T, CADD 18.20
- K9R (p.Lys9Arg), rs2465679456, ClinGen CA346601216, ClinVar RCV003112608, Uncertain significance, Hereditary spastic paraplegia 4
- K9N (p.Lys9Asn), gnomAD 2-32063858-G-C, REVEL 0.22, CADD 22.20
- K9K (p.Lys9Lys), rs1445410182, gnomAD 2-32063858-G-A, CADD 13.60
- K10R (p.Lys10Arg), rs2148685090, ClinGen CA346601224, ClinVar RCV001762930, Ensembl rs2148685090, REVEL 0.37, CADD 24.30, Uncertain significance, not provided
- K10N (p.Lys10Asn), gnomAD 2-32063861-G-C, REVEL 0.38, CADD 26.70
- K10K (p.Lys10Lys), rs768928614, gnomAD 2-32063861-G-A, CADD 13.90
- K11R (p.Lys11Arg), TOPMed rs1201815863, gnomAD rs1201815863, REVEL 0.25, CADD 24.00
- K11del (p.Lys11del), gnomAD 2-32063854-GGAA-G, CADD 21.00
- K11E (p.Lys11Glu), gnomAD 2-32063862-A-G, REVEL 0.36, CADD 24.30
- K11K (p.Lys11Lys), gnomAD 2-32063864-A-G, CADD 15.20
- G12S (p.Gly12Ser), rs2465679498, ClinGen CA346601236, ClinVar RCV002717827, REVEL 0.34, CADD 23.20, Uncertain significance, Inborn genetic diseases
- G12C (p.Gly12Cys), gnomAD 2-32063865-G-T, REVEL 0.47, CADD 28.40
- G12V (p.Gly12Val), gnomAD 2-32063866-G-T, REVEL 0.43, CADD 24.10
- G12D (p.Gly12Asp), gnomAD 2-32063866-G-A, REVEL 0.43, CADD 22.90
- G12G (p.Gly12Gly), gnomAD 2-32063867-C-A, CADD 14.40
- S13A (p.Ser13Ala), ExAC rs781222498, TOPMed rs781222498, gnomAD rs781222498, REVEL 0.33, CADD 19.40, Likely benign
- S13P (p.Ser13Pro), ExAC rs781222498, TOPMed rs781222498, gnomAD rs781222498, REVEL 0.29, CADD 23.00, Likely benign
- S13T (p.Ser13Thr), rs781222498, ClinGen CA1600460, ClinVar RCV001903520, ClinVar RCV002473320, REVEL 0.27, CADD 22.00, Conflicting interpretations, not provided; Hereditary spastic paraplegia 4
- S13Y (p.Ser13Tyr), gnomAD 2-32063869-C-A, REVEL 0.28, CADD 20.90
- S13S (p.Ser13Ser), rs769680370, gnomAD 2-32063870-C-T, CADD 14.20
- G14S (p.Gly14Ser), rs2465679591, ClinGen CA346601246, ClinVar RCV002975576, REVEL 0.29, CADD 23.10, Uncertain significance, Hereditary spastic paraplegia 4
- G14C (p.Gly14Cys), gnomAD 2-32063871-G-T, REVEL 0.31, CADD 28.50
- G14D (p.Gly14Asp), gnomAD 2-32063872-G-A, REVEL 0.34, CADD 23.90
- G14G (p.Gly14Gly), gnomAD 2-32063873-C-A, CADD 13.30
- G15D (p.Gly15Asp), gnomAD rs1330833579, REVEL 0.25, CADD 22.10
- G15R (p.Gly15Arg), gnomAD rs1319401583, REVEL 0.32, CADD 24.50
- G15S (p.Gly15Ser), gnomAD rs1319401583, REVEL 0.26, CADD 20.50, Uncertain significance, Hereditary spastic paraplegia 4
- G15C (p.Gly15Cys), gnomAD 2-32063874-G-T, REVEL 0.34, CADD 23.60
- G15V (p.Gly15Val), gnomAD 2-32063875-G-T, REVEL 0.29, CADD 22.10
- G15G (p.Gly15Gly), rs1221944437, gnomAD 2-32063876-C-T, CADD 14.40
- A16P (p.Ala16Pro), ExAC rs773348749, TOPMed rs773348749, gnomAD rs773348749, REVEL 0.33, CADD 14.30
- A16T (p.Ala16Thr), ExAC rs773348749, TOPMed rs773348749, gnomAD rs773348749, REVEL 0.33, CADD 17.90, Uncertain significance, Inborn genetic diseases
- A16V (p.Ala16Val), ExAC rs770931525, gnomAD rs770931525, REVEL 0.28, CADD 22.60
- A16S (p.Ala16Ser), gnomAD 2-32063877-G-T, REVEL 0.35, CADD 11.00
- A16G (p.Ala16Gly), gnomAD 2-32063878-C-G, REVEL 0.26, CADD 19.40
- A16D (p.Ala16Asp), gnomAD 2-32063878-C-A, REVEL 0.28, CADD 22.60
- A16A (p.Ala16Ala), gnomAD 2-32063879-C-A, CADD 14.00
- S17N (p.Ser17Asn), Ensembl rs1676386884, REVEL 0.28, CADD 23.60
- S17R (p.Ser17Arg), rs1303074496, ClinGen CA346601267, ClinVar RCV001936355, TOPMed rs1303074496, REVEL 0.21, CADD 21.10, Likely benign, Hereditary spastic paraplegia 4
- S17G (p.Ser17Gly), gnomAD 2-32063880-A-G, REVEL 0.29, CADD 19.00
- S17I (p.Ser17Ile), gnomAD 2-32063881-G-T, REVEL 0.27, CADD 24.10
- S17S (p.Ser17Ser), gnomAD 2-32063882-C-T, CADD 14.80
- N18I (p.Asn18Ile), Ensembl rs1676387120, REVEL 0.32, CADD 23.10
- N18T (p.Asn18Thr), Ensembl rs1676387120
- N18K (p.Asn18Lys), gnomAD 2-32063885-C-A, REVEL 0.23, CADD 21.80
- N18N (p.Asn18Asn), rs1558605352, gnomAD 2-32063885-C-T, CADD 13.60
- P19A (p.Pro19Ala), rs372349942, ClinGen CA346601276, ClinVar RCV004798943, AlphaMissense 0.08, MetaLR 0.54, Likely pathogenic, Hereditary spastic paraplegia 4
- P19L (p.Pro19Leu), Ensembl rs1474477736, REVEL 0.26, CADD 23.70, Uncertain significance, Inborn genetic diseases
- P19R (p.Pro19Arg), Ensembl rs1474477736, Uncertain significance, not provided
- P19S (p.Pro19Ser), rs372349942, ClinGen CA10615118, ClinVar RCV000317684, ClinVar RCV004767235, REVEL 0.28, AlphaMissense 0.08, Uncertain significance, not specified; Hereditary spastic paraplegia 4
- P19T (p.Pro19Thr), ExAC rs372349942, TOPMed rs372349942, gnomAD rs372349942, REVEL 0.27, AlphaMissense 0.08, Uncertain significance
- P19del (p.Pro19del), rs778861675, gnomAD 2-32063885-CCCG-C, CADD 20.30
- P19Q (p.Pro19Gln), gnomAD 2-32063887-C-A, REVEL 0.32, CADD 24.50
- P19P (p.Pro19Pro), gnomAD 2-32063888-G-A, CADD 14.90
- V20D (p.Val20Asp), rs2465679807, ClinGen CA2580066368, ClinVar RCV002511959, Pathogenic
- V20L (p.Val20Leu), Ensembl rs931391628, REVEL 0.28, CADD 22.00, Uncertain significance, not provided
- V20M (p.Val20Met), gnomAD 2-32063889-G-A, REVEL 0.31, CADD 22.70
- V20A (p.Val20Ala), gnomAD 2-32063890-T-C, REVEL 0.30, CADD 18.40
- V20V (p.Val20Val), rs752272987, gnomAD 2-32063891-G-T, CADD 13.70
- P21L (p.Pro21Leu), TOPMed rs1305710044, gnomAD rs1305710044, REVEL 0.28, CADD 22.80
- P21T (p.Pro21Thr), Ensembl rs865867577, REVEL 0.29, CADD 21.90
- P21H (p.Pro21His), gnomAD 2-32063893-C-A, REVEL 0.28, CADD 23.60
- P21P (p.Pro21Pro), rs1676388360, gnomAD 2-32063894-T-C, CADD 15.10
- P22A (p.Pro22Ala), rs762209469, ClinGen CA1600472, ClinVar RCV000863622, ClinVar RCV003243356, REVEL 0.25, CADD 14.90, Likely benign, Inborn genetic diseases; Hereditary spastic paraplegia 4
- P22S (p.Pro22Ser), ExAC rs762209469, TOPMed rs762209469, gnomAD rs762209469, REVEL 0.23, CADD 18.90, Likely benign, Inborn genetic diseases
- P22T (p.Pro22Thr), gnomAD 2-32063895-C-A, REVEL 0.24, CADD 19.30
- P22P (p.Pro22Pro), rs1262209200, gnomAD 2-32063897-C-T, CADD 14.90
- R23G (p.Arg23Gly), rs2465679891, ClinGen CA346601294, ClinVar RCV002996475, REVEL 0.34, CADD 22.70, Uncertain significance, Hereditary spastic paraplegia 4
- R23K (p.Arg23Lys), rs558882317, ClinGen CA1600473, ClinVar RCV000842632, ClinVar RCV001521667, REVEL 0.26, CADD 20.10, Benign/Likely benign, Hereditary spastic paraplegia; Hereditary spastic paraplegia 4; not provided
- R23S (p.Arg23Ser), TOPMed rs1676389249
- R23T (p.Arg23Thr), gnomAD 2-32063899-G-C, REVEL 0.26, CADD 22.60
- R23M (p.Arg23Met), gnomAD 2-32063899-G-T, REVEL 0.37, CADD 23.10
- R23R (p.Arg23Arg), gnomAD 2-32063900-G-A, CADD 15.20
- P24S (p.Pro24Ser), rs2465679933, ClinGen CA346601302, ClinVar RCV002740369, REVEL 0.23, CADD 22.40, Uncertain significance, Hereditary spastic paraplegia 4
- P24T (p.Pro24Thr), gnomAD 2-32063901-C-A, REVEL 0.24, CADD 23.10
- P24H (p.Pro24His), gnomAD 2-32063902-C-A, REVEL 0.30, CADD 23.40
- P24P (p.Pro24Pro), gnomAD 2-32063903-T-G, CADD 16.00
- P25A (p.Pro25Ala), rs758920536, ClinGen CA346601307, ClinVar RCV002577227, ClinVar RCV002577228, REVEL 0.31, CADD 19.80, Conflicting interpretations, Inborn genetic diseases; Hereditary spastic paraplegia 4
- P25L (p.Pro25Leu), Ensembl rs1573026974, REVEL 0.37, CADD 22.90, Uncertain significance, Hereditary spastic paraplegia 4
- P25S (p.Pro25Ser), rs758920536, ClinGen CA1600474, ClinVar RCV002474440, ExAC rs758920536, REVEL 0.29, CADD 22.30, Uncertain significance, not provided
- P25Q (p.Pro25Gln), gnomAD 2-32063905-C-A, REVEL 0.35, CADD 22.60
- P25P (p.Pro25Pro), rs926267776, gnomAD 2-32063906-G-A, CADD 15.10
- P26A (p.Pro26Ala), ExAC rs780359337, gnomAD rs780359337
- P26S (p.Pro26Ser), ExAC rs780359337, gnomAD rs780359337, REVEL 0.33, CADD 21.10
- P26P (p.Pro26Pro), rs572109743, gnomAD 2-32063909-C-A, CADD 13.60
- P27L (p.Pro27Leu), rs1361493550, ClinGen CA346601321, cosmic curated COSV10453, ClinVar RCV001066648, REVEL 0.21, CADD 22.30, Uncertain significance, Inborn genetic diseases; Hereditary spastic paraplegia 4
- P27S (p.Pro27Ser), cosmic curated COSV10645, TOPMed rs1325448402, gnomAD rs1325448402
- P27T (p.Pro27Thr), TOPMed rs1325448402, gnomAD rs1325448402, Uncertain significance, Hereditary spastic paraplegia 4
- p.Pro27 Pro42del, rs2148685190, gnomAD 2-32063900-GCCTCC, CADD 20.10
- P27R (p.Pro27Arg), gnomAD 2-32063911-C-G, REVEL 0.21, CADD 21.20
- P27P (p.Pro27Pro), rs2148685236, gnomAD 2-32063912-T-C, CADD 12.80
- C28G (p.Cys28Gly), Ensembl rs2148685246
- C28S (p.Cys28Ser), rs1676390484, ClinGen CA346601326, ClinVar RCV001238954, TOPMed rs1676390484, REVEL 0.20, CADD 17.40, Uncertain significance, Hereditary spastic paraplegia 4
- C28W (p.Cys28Trp), Ensembl rs2148685255, REVEL 0.26, CADD 23.30
- C28Y (p.Cys28Tyr), gnomAD 2-32063914-G-A, REVEL 0.17, CADD 21.60
- C28F (p.Cys28Phe), gnomAD 2-32063914-G-T, REVEL 0.17, CADD 21.70
- L29P (p.Leu29Pro), Ensembl rs1676390679, REVEL 0.32, CADD 14.30
- L29Q (p.Leu29Gln), Ensembl rs1676390679
- L29R (p.Leu29Arg), Ensembl rs1676390679
- L29V (p.Leu29Val), TOPMed rs1676390571, REVEL 0.17, CADD 5.83
- L29L (p.Leu29Leu), rs1373511876, gnomAD 2-32063918-G-T, CADD 13.20
- A30G (p.Ala30Gly), ExAC rs781516235, TOPMed rs781516235, gnomAD rs781516235, REVEL 0.20, CADD 15.40, Likely benign
- A30S (p.Ala30Ser), gnomAD rs1676390895, REVEL 0.17, CADD 17.60
- A30V (p.Ala30Val), rs781516235, ClinGen CA1600478, ClinVar RCV000814318, ExAC rs781516235, REVEL 0.17, CADD 16.00, Likely benign, Hereditary spastic paraplegia 4
- A30D (p.Ala30Asp), gnomAD 2-32063920-C-A, REVEL 0.19, CADD 16.10
- A30A (p.Ala30Ala), gnomAD 2-32063921-C-T, CADD 13.30
- P31L (p.Pro31Leu), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10018, REVEL 0.21, CADD 22.00, Variant assessed as somatic; moderate impact.
- P31S (p.Pro31Ser), gnomAD 2-32063922-C-T, REVEL 0.28, CADD 8.24
- P31H (p.Pro31His), gnomAD 2-32063923-C-A, REVEL 0.25, CADD 21.70
- P31P (p.Pro31Pro), rs748312175, gnomAD 2-32063924-C-A, CADD 14.20
- A32P (p.Ala32Pro), cosmic curated COSV10965, gnomAD rs1676391613, REVEL 0.36, CADD 22.20, Uncertain significance, not provided
- A32T (p.Ala32Thr), gnomAD rs1676391613, REVEL 0.19, CADD 21.50
- A32R (p.Ala32Arg), rs1676391139, gnomAD 2-32063919-G-GC, CADD 26.50
- A32V (p.Ala32Val), gnomAD 2-32063926-C-T, REVEL 0.20, CADD 20.90
- A32A (p.Ala32Ala), rs200837566, gnomAD 2-32063927-C-T, CADD 14.90
- P33A (p.Pro33Ala), rs1403480959, ClinGen CA346601353, ClinVar RCV002263201, ClinVar RCV003633607, REVEL 0.23, CADD 18.60, Conflicting interpretations, Hereditary spastic paraplegia 4; not provided
- P33L (p.Pro33Leu), rs777721232, ClinGen CA1600482, cosmic curated COSV10582, ClinVar RCV000424827, REVEL 0.22, CADD 22.20, Uncertain significance, Hereditary spastic paraplegia 4; not provided
- P33S (p.Pro33Ser), rs1403480959, ClinGen CA346601354, ClinVar RCV003112961, TOPMed rs1403480959, REVEL 0.23, CADD 21.00, Uncertain significance, Hereditary spastic paraplegia 4
- p.Pro33 Ala35del, rs745951969, gnomAD 2-32063921-CCCCGC, CADD 19.60
- P33T (p.Pro33Thr), gnomAD 2-32063928-C-A, REVEL 0.26, CADD 19.90
- P33P (p.Pro33Pro), rs1573027124, gnomAD 2-32063930-T-C, CADD 13.10
- P34L (p.Pro34Leu), rs771019519, ClinGen CA1600484, ClinVar RCV001342255, ExAC rs771019519, REVEL 0.18, CADD 21.60, Uncertain significance, Hereditary spastic paraplegia 4
- P34S (p.Pro34Ser), ExAC rs749021726, TOPMed rs749021726, gnomAD rs749021726, REVEL 0.19, CADD 20.00, Uncertain significance, Hereditary spastic paraplegia 4
- P34T (p.Pro34Thr), rs749021726, ClinGen CA1600483, ClinVar RCV003634241, ExAC rs749021726, REVEL 0.16, CADD 18.40, Likely benign, Hereditary spastic paraplegia 4
- P34A (p.Pro34Ala), gnomAD 2-32063931-C-G, REVEL 0.26, CADD 16.40
- P34P (p.Pro34Pro), rs1304986567, gnomAD 2-32063933-C-T, CADD 14.20
- A35P (p.Ala35Pro), 1000Genomes rs560002466, ExAC rs560002466, gnomAD rs560002466, REVEL 0.32, CADD 22.70
- A35S (p.Ala35Ser), 1000Genomes rs560002466, ExAC rs560002466, gnomAD rs560002466, REVEL 0.22, CADD 19.40
- A35T (p.Ala35Thr), gnomAD 2-32063934-G-A, REVEL 0.21, CADD 21.90
- A35V (p.Ala35Val), gnomAD 2-32063935-C-T, REVEL 0.20, CADD 20.00
- A35A (p.Ala35Ala), gnomAD 2-32063936-C-T, CADD 14.10
- A36P (p.Ala36Pro), TOPMed rs1482010474, gnomAD rs1482010474, REVEL 0.28, CADD 20.90
- A36S (p.Ala36Ser), TOPMed rs1482010474, gnomAD rs1482010474
- A36T (p.Ala36Thr), TOPMed rs1482010474, gnomAD rs1482010474, REVEL 0.18, CADD 21.40
- A36A (p.Ala36Ala), rs1261214882, gnomAD 2-32063939-C-T, CADD 13.90
- G37E (p.Gly37Glu), NCI-TCGA TCGA novel, REVEL 0.31, CADD 15.00, Variant assessed as somatic; moderate impact.
- G37R (p.Gly37Arg), rs771455657, ClinGen CA1600487, NCI-TCGA Cosmic COSV1001, cosmic curated COSV10018, REVEL 0.28, CADD 17.60, Conflicting interpretations, not provided; Hereditary spastic paraplegia 4
- G37W (p.Gly37Trp), rs771455657, ClinGen CA346601373, cosmic curated COSV59518, ClinVar RCV001391567, REVEL 0.31, CADD 23.20, Uncertain significance, Spastic paraplegia
- P38A (p.Pro38Ala), gnomAD rs1219971550, REVEL 0.27, CADD 16.00
- P38L (p.Pro38Leu), rs1041662261, ClinGen CA346601380, ClinVar RCV001141199, TOPMed rs1041662261, REVEL 0.29, CADD 15.90, Uncertain significance, Hereditary spastic paraplegia 4
- P38R (p.Pro38Arg), rs1041662261, ClinGen CA16610961, ClinVar RCV000464226, ClinVar RCV004668985, REVEL 0.24, CADD 14.80, Uncertain significance, Hereditary spastic paraplegia 4; Inborn genetic diseases
- P38S (p.Pro38Ser), gnomAD 2-32063943-C-T, REVEL 0.26, CADD 17.90
- P38P (p.Pro38Pro), gnomAD 2-32063945-G-A, CADD 12.20
- A39D (p.Ala39Asp), rs1176214835, ClinGen CA346601385, ClinVar RCV002661693, ClinVar RCV006560816, REVEL 0.32, CADD 17.80, Uncertain significance, not provided; Inborn genetic diseases
- A39T (p.Ala39Thr), TOPMed rs1676394003, gnomAD rs1676394003, REVEL 0.24, CADD 20.70, Uncertain significance, Hereditary spastic paraplegia 4
- A39A (p.Ala39Ala), rs760308500, gnomAD 2-32063948-C-G, CADD 11.70
- P40L (p.Pro40Leu), rs1183243810, ClinGen CA346601390, ClinVar RCV002970878, TOPMed rs1183243810, REVEL 0.25, CADD 18.30, Likely benign, Hereditary spastic paraplegia 4
Public SPAST analysis runs
- SPAST analysis run — SPAST (1,384 variants) — completed 2026-08-22