IDS (Iduronate 2-sulfatase) variants and mutations
IDS (also known as Iduronate 2-sulfatase) is a human protein-coding gene encoding an iduronate 2-sulfatase protein. It removes sulfate groups from iduronate-containing glycosaminoglycans during lysosomal degradation. Loss-of-function variants cause X-linked Hunter syndrome, with progressive accumulation of dermatan and heparan sulfate affecting multiple organs and, in severe disease, the nervous system. This analysis covers 897 IDS variants and mutations. Of these, 71% have computational variant effect predictions. Disease context includes mucopolysaccharidosis type 2, hereditary disease, and mucopolysaccharidosis. Example IDS variants include M1T, P2T, and P3L.
Variant analysis overview
- Gene: IDS
- Protein: Iduronate 2-sulfatase
- UniProt accession: P22304
- Organism: Homo sapiens
- Variants analyzed: 897
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 691 unspecified-consequence records; 98 synonymous variants; 93 missense variants; 1 stop-gained variants; 3 frameshift variants; 2 in-frame insertions; 2 stop lost; 1 splice-region variants; 6 substitution
- Prediction scores: 641 variants have prediction scores (71% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: mucopolysaccharidosis type 2, hereditary disease, mucopolysaccharidosis, mucopolysaccharidosis type 2, severe form, mucopolysaccharidosis type 3A, mucopolysaccharidosis type 2, attenuated form, epidermolysis bullosa simplex with nail dystrophy, cranioectodermal dysplasia, 3M syndrome, mandibuloacral dysplasia, osteogenesis imperfecta, Torg-Winchester syndrome.
Protein structure and variant hotspots
- Protein features: 5 binding sites; 8 post-translational modification sites.
- PTM context: 10 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable IDS variants
Examples include M1T, P2T, P3L, P4L, P4R, P4T, R5G, R5L. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1T (p.Met1Thr), rs2124069617, ClinGen CA414528847, ClinVar RCV001965495, MetaLR 0.92, MetaSVM 0.76, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- P2T (p.Pro2Thr), TOPMed rs1382230677, gnomAD rs1382230677, REVEL 0.29, CADD 6.93, Pathogenic, Mucopolysaccharidosis, MPS-II
- P3L (p.Pro3Leu), Ensembl rs2089516652
- P4L (p.Pro4Leu), gnomAD rs1557340625, REVEL 0.37, CADD 15.80
- P4R (p.Pro4Arg), gnomAD rs1557340625
- P4T (p.Pro4Thr), rs2520911157, ClinGen CA414528778, ClinVar RCV002893595, Uncertain significance, Inborn genetic diseases
- R5G (p.Arg5Gly), ESP rs141900718, ExAC rs141900718, TOPMed rs141900718, gnomAD rs141900718, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II; Inborn genetic diseases
- R5L (p.Arg5Leu), NCI-TCGA TCGA novel, REVEL 0.37, CADD 6.99, Variant assessed as somatic; moderate impact.
- R5W (p.Arg5Trp), rs141900718, ClinGen CA10537765, ClinVar RCV002175566, ESP rs141900718, REVEL 0.46, CADD 10.90, Benign, Mucopolysaccharidosis, MPS-II
- G7R (p.Gly7Arg), TOPMed rs1052659546, gnomAD rs1052659546, REVEL 0.39, CADD 13.60
- R8* (p.Arg8Ter), rs1602750610, ClinGen CA414528693, ClinVar RCV001216081, TOPMed rs1602750610, Pathogenic
- R8L (p.Arg8Leu), rs782621858, ClinGen CA10537762, ClinVar RCV000934628, ClinVar RCV002427322, REVEL 0.29, CADD 6.88, Benign/Likely benign, Inborn genetic diseases; not provided; Mucopolysaccharidosis, MPS-II
- R8P (p.Arg8Pro), ExAC rs782621858, TOPMed rs782621858, gnomAD rs782621858, Benign
- R8Q (p.Arg8Gln), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, Variant assessed as somatic; moderate impact.
- G9C (p.Gly9Cys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G9S (p.Gly9Ser), rs1557340605, gnomAD rs1557340605, REVEL 0.35, CADD 4.88, Variant assessed as somatic; moderate impact.
- L10F (p.Leu10Phe), rs2067278577, ClinGen CA414528648, ClinVar RCV002939215, ClinVar RCV003621677, REVEL 0.38, CADD 9.12, Conflicting interpretations, Inborn genetic diseases; Mucopolysaccharidosis, MPS-II
- L11F (p.Leu11Phe), rs1557340600, ClinGen CA414528622, ClinVar RCV003832530, ClinVar RCV005856576, REVEL 0.30, CADD 8.41, Conflicting interpretations, Inborn genetic diseases; Mucopolysaccharidosis, MPS-II
- L11I (p.Leu11Ile), gnomAD rs1557340600, REVEL 0.24, CADD 8.15, Likely benign
- W12* (p.Trp12Ter), rs2520910742, ClinGen CA414528590, ClinVar RCV003509092, CADD 32.00, Pathogenic
- W12R (p.Trp12Arg), rs1557340598, ClinGen CA414528609, ClinVar RCV002008110, gnomAD rs1557340598, REVEL 0.54, CADD 8.14, Likely benign, Mucopolysaccharidosis, MPS-II
- G14D (p.Gly14Asp), rs373389352, ClinGen CA10537758, ClinVar RCV001519863, ClinVar RCV001826378, REVEL 0.56, CADD 12.90, Benign/Likely benign, Inborn genetic diseases; Mucopolysaccharidosis, MPS-II
- G14R (p.Gly14Arg), gnomAD rs1557340590, REVEL 0.52, CADD 8.38
- G14S (p.Gly14Ser), gnomAD rs1557340590
- V16F (p.Val16Phe), Ensembl rs2089515649
- L17V (p.Leu17Val), ExAC rs781834400, TOPMed rs781834400, gnomAD rs781834400, REVEL 0.35, CADD 10.10, Likely benign
- S18R (p.Ser18Arg), ExAC rs782607292, TOPMed rs782607292, gnomAD rs782607292, REVEL 0.57, CADD 8.79, Likely benign
- S19Y (p.Ser19Tyr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V20I (p.Val20Ile), ESP rs11549010, ExAC rs11549010, TOPMed rs11549010, gnomAD rs11549010, REVEL 0.16, CADD 0.11, Likely benign
- V20L (p.Val20Leu), rs11549010, ClinGen CA10537755, ClinVar RCV002995901, ClinVar RCV002995902, REVEL 0.29, CADD 0.17, Conflicting interpretations, Inborn genetic diseases; Mucopolysaccharidosis, MPS-II
- C21* (p.Cys21Ter), NCI-TCGA Cosmic COSV6171, cosmic curated COSV61712, CADD 24.30, Variant assessed as somatic; high impact.
- V22D (p.Val22Asp), gnomAD rs1557340581, REVEL 0.60, CADD 10.00
- V22I (p.Val22Ile), rs2520910307, ClinGen CA414528356, ClinVar RCV003090619, REVEL 0.23, CADD 0.08, Uncertain significance, Mucopolysaccharidosis, MPS-II
- A23T (p.Ala23Thr), rs782815584, NCI-TCGA Cosmic COSV6171, cosmic curated COSV61711, ExAC rs782815584, REVEL 0.31, CADD 3.04, Uncertain significance, Mucopolysaccharidosis, MPS-III-A
- S26A (p.Ser26Ala), TOPMed rs2089514984
- S26C (p.Ser26Cys), rs1557340575, NCI-TCGA Cosmic COSV6171, cosmic curated COSV61715, gnomAD rs1557340575, REVEL 0.43, CADD 8.32, Variant assessed as somatic; moderate impact.
- E27K (p.Glu27Lys), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, NCI-TCGA Cosmic COSV6171, Variant assessed as somatic; moderate impact.
- T28R (p.Thr28Arg), NCI-TCGA TCGA novel, REVEL 0.39, CADD 1.44, Variant assessed as somatic; moderate impact.
- Q29K (p.Gln29Lys), gnomAD rs1557340571, REVEL 0.41, CADD 8.85
- Q29L (p.Gln29Leu), TOPMed rs1253381041, REVEL 0.33, CADD 3.58, Uncertain significance, Mucopolysaccharidosis, MPS-II
- A30V (p.Ala30Val), gnomAD rs2089514573, REVEL 0.29, CADD 8.67
- N31S (p.Asn31Ser), rs184190241, ClinGen CA337036768, ClinVar RCV002648227, 1000Genomes rs184190241, REVEL 0.23, CADD 0.71, Likely benign, Mucopolysaccharidosis, MPS-II
- T33I (p.Thr33Ile), rs1557340562, ClinGen CA414528138, ClinVar RCV003622337, TOPMed rs1557340562, REVEL 0.32, CADD 10.00, Uncertain significance, Mucopolysaccharidosis, MPS-II
- T33S (p.Thr33Ser), rs782158763, ClinGen CA10537750, ClinVar RCV001279580, 1000Genomes rs782158763, REVEL 0.31, CADD 0.15, Likely benign, Mucopolysaccharidosis, MPS-II
- T34A (p.Thr34Ala), rs2520909700, ClinGen CA414528131, ClinVar RCV002306163, NCI-TCGA TCGA novel, Uncertain significance, not provided
- T34I (p.Thr34Ile), rs1156672457, ClinGen CA414528121, ClinVar RCV002464930, TOPMed rs1156672457, REVEL 0.34, CADD 21.20, Uncertain significance, not provided
- T34K (p.Thr34Lys), rs1156672457, ClinGen CA414528125, ClinVar RCV003822459, REVEL 0.43, CADD 12.90, Uncertain significance, Mucopolysaccharidosis, MPS-II
- D35G (p.Asp35Gly), rs144081417, ClinGen CA241305, ClinVar RCV000675884, ClinVar RCV001081199, REVEL 0.42, CADD 14.30, Benign
- D35H (p.Asp35His), rs2089514224, ClinGen CA414528115, ClinVar RCV001290989, ClinVar RCV004793370, AlphaMissense 0.09, MetaLR 0.95, Likely pathogenic, not provided; Mucopolysaccharidosis, MPS-II
- D35V (p.Asp35Val), rs144081417, ClinGen CA414527975, ClinVar RCV002269412, ESP rs144081417, REVEL 0.42, CADD 16.60, Uncertain significance, not provided
- A36S (p.Ala36Ser), rs782736039, ExAC rs782736039, TOPMed rs782736039, gnomAD rs782736039, REVEL 0.38, CADD 0.66, Uncertain significance
- A36T (p.Ala36Thr), rs782736039, ClinGen CA10537733, ClinVar RCV002584529, ExAC rs782736039, REVEL 0.37, CADD 2.82, Uncertain significance, Mucopolysaccharidosis, MPS-II
- N38K (p.Asn38Lys), ESP rs149512799, ExAC rs149512799, TOPMed rs149512799, gnomAD rs149512799, REVEL 0.80, CADD 18.30, Likely benign
- V39D (p.Val39Asp), rs2520902410, ClinGen CA414527906, ClinVar RCV003131209, Uncertain significance, Mucopolysaccharidosis, MPS-II
- V39I (p.Val39Ile), rs931984538, ClinVar RCV004593515, TOPMed rs931984538, gnomAD rs931984538, REVEL 0.40, CADD 12.20, Uncertain significance, not provided
- L40P (p.Leu40Pro), rs2520902336, ClinGen CA414527890, ClinVar RCV003135719, Uncertain significance, Mucopolysaccharidosis, MPS-II
- L41I (p.Leu41Ile), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, Ensembl rs2089505355, Variant assessed as somatic; moderate impact., in MPS2
- L41P (p.Leu41Pro), UniProt VAR 026915, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- L41R (p.Leu41Arg), Ensembl rs2089505287, REVEL 0.87, CADD 24.40
- I42M (p.Ile42Met), 1000Genomes rs146963087, ESP rs146963087, ExAC rs146963087, TOPMed rs146963087, Uncertain significance, not specified
- I42V (p.Ile42Val), rs2089505177, ClinGen CA414527865, ClinVar RCV001040147, Ensembl rs2089505177, AlphaMissense 0.11, MetaLR 0.99, Uncertain significance, Mucopolysaccharidosis, MPS-II
- V44L (p.Val44Leu), TOPMed rs1308426956, gnomAD rs1308426956
- V44M (p.Val44Met), rs1308426956, TOPMed rs1308426956, gnomAD rs1308426956, REVEL 0.75, CADD 24.20, Variant assessed as somatic; moderate impact.
- D45G (p.Asp45Gly), rs2520901934, ClinGen CA414527795, ClinVar RCV003222542, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- D45H (p.Asp45His), rs869025301, ClinGen CA356953, ClinVar RCV000207419, Ensembl rs869025301, AlphaMissense 0.96, MetaLR 1.00, Pathogenic, in MPS2
- D45N (p.Asp45Asn), rs869025301, UniProt VAR 007313, Ensembl rs869025301, AlphaMissense 0.96, MetaLR 1.00, Pathogenic, Mucopolysaccharidosis, MPS-II
- D46E (p.Asp46Glu), rs2520901887, ClinGen CA414527767, ClinVar RCV003447459, Pathogenic, Mucopolysaccharidosis, MPS-II
- D46N (p.Asp46Asn), rs2089504816, ClinGen CA414527783, NCI-TCGA Cosmic COSV6171, cosmic curated COSV61714, AlphaMissense 0.96, MetaLR 1.00, Pathogenic, Mucopolysaccharidosis, MPS-II
- D46Y (p.Asp46Tyr), rs2089504816, ClinGen CA414527779, ClinVar RCV001290992, Ensembl rs2089504816, REVEL 0.99, AlphaMissense 0.96, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- R48C (p.Arg48Cys), rs1412895796, ClinGen CA414527742, NCI-TCGA Cosmic COSV6171, cosmic curated COSV61712, AlphaMissense 0.47, MetaLR 1.00, Conflicting interpretations, not specified; Mucopolysaccharidosis, MPS-II
- R48H (p.Arg48His), NCI-TCGA Cosmic COSV6171, cosmic curated COSV61711, REVEL 0.96, CADD 26.80, Uncertain significance, Mucopolysaccharidosis, MPS-II
- R48P (p.Arg48Pro), rs1569560528, ClinGen CA414527737, ClinVar RCV000780348, UniProt VAR 007314, AlphaMissense 0.95, MetaLR 1.00, Pathogenic, Mucopolysaccharidosis, MPS-II
- P49L (p.Pro49Leu), TOPMed rs1335589314, gnomAD rs1335589314, REVEL 0.84, CADD 24.90
- Y54* (p.Tyr54Ter), rs141088021, ClinGen CA414527636, ClinVar RCV001291746, 1000Genomes rs141088021, Pathogenic, in MPS2
- Y54D (p.Tyr54Asp), UniProt VAR 007315, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- G55V (p.Gly55Val), rs2520901561, ClinGen CA414527616, ClinVar RCV002902634, Uncertain significance, Inborn genetic diseases
- D56N (p.Asp56Asn), rs781919816, ClinGen CA414527612, ClinVar RCV002574982, AlphaMissense 0.20, MetaLR 0.98, Uncertain significance, Mucopolysaccharidosis, MPS-II
- D56Y (p.Asp56Tyr), ExAC rs781919816, REVEL 0.69, AlphaMissense 0.20, Likely benign, not provided
- V59L (p.Val59Leu), NCI-TCGA TCGA novel, REVEL 0.41, CADD 9.12, Variant assessed as somatic; moderate impact.
- V59M (p.Val59Met), gnomAD rs1557340410
- R60K (p.Arg60Lys), TOPMed rs2089504337, gnomAD rs2089504337, REVEL 0.42, CADD 12.80
- R60M (p.Arg60Met), TOPMed rs2089504337, gnomAD rs2089504337, REVEL 0.59, CADD 19.10
- S61F (p.Ser61Phe), rs2124065955, ClinGen CA414527509, ClinVar RCV001376698, Ensembl rs2124065955, AlphaMissense 0.87, MetaLR 1.00, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- S61P (p.Ser61Pro), rs113993955, ClinGen CA350785, ClinVar RCV000206790, ClinVar RCV001092169, AlphaMissense 0.86, MetaLR 0.99, Pathogenic
- P62A (p.Pro62Ala), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, Variant assessed as somatic; moderate impact.
- N63D (p.Asn63Asp), rs193302909, ClinGen CA337036725, ClinVar RCV000790544, UniProt VAR 007316, AlphaMissense 0.71, MetaLR 1.00, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- I64N (p.Ile64Asn), rs781997631, ClinGen CA350641, ClinVar RCV000206626, ExAC rs781997631, AlphaMissense 0.89, MetaLR 0.98, Pathogenic
- I64T (p.Ile64Thr), ExAC rs781997631, gnomAD rs781997631, REVEL 0.95, AlphaMissense 0.89, Uncertain significance, Inborn genetic diseases; not specified
- Q66* (p.Gln66Ter), rs1557340403, ClinGen CA414527410, ClinVar RCV000625940, Ensembl rs1557340403, Pathogenic
- Q66R (p.Gln66Arg), ExAC rs782375828, TOPMed rs782375828, gnomAD rs782375828, REVEL 0.63, CADD 21.60
- L67M (p.Leu67Met), rs2520901163, ClinGen CA414527392, ClinVar RCV002417062, Uncertain significance, Inborn genetic diseases
- L67P (p.Leu67Pro), rs2520901143, ClinGen CA414527386, ClinVar RCV003135716, Conflicting interpretations, Mucopolysaccharidosis, MPS-II
- A68E (p.Ala68Glu), UniProt VAR 007317, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- S69* (p.Ser69Ter), rs2124065847, ClinGen CA2499226402, ClinVar RCV001375631, Ensembl rs2124065847, Pathogenic
- S69T (p.Ser69Thr), gnomAD rs1557340397, REVEL 0.61, CADD 22.50, Likely benign, Mucopolysaccharidosis, MPS-II
- H70Y (p.His70Tyr), gnomAD rs1557340393
- H70PfsX29, rs797044671, Pathogenic
- S71I (p.Ser71Ile), rs113993954, ClinGen CA414527310, ClinVar RCV001553790, Ensembl rs113993954, AlphaMissense 0.88, MetaLR 1.00, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- S71N (p.Ser71Asn), rs113993954, ClinGen CA337036723, cosmic curated COSV61714, ClinVar RCV001912365, AlphaMissense 0.88, MetaLR 1.00, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- S71R (p.Ser71Arg), rs2520900915, ClinGen CA414527303, ClinVar RCV002430502, ClinVar RCV004596551, Likely pathogenic, Inborn genetic diseases; Mucopolysaccharidosis, MPS-II
- L72R (p.Leu72Arg), gnomAD rs2089503838, REVEL 0.67, CADD 22.80
- L73F (p.Leu73Phe), UniProt VAR 026917, Uncertain significance, Mucopolysaccharidosis, MPS-II
- Q75* (p.Gln75Ter), rs2089503778, ClinGen CA414527234, ClinVar RCV001291749, Ensembl rs2089503778, Pathogenic
- Q75E (p.Gln75Glu), rs2089503778, ClinGen CA414527237, ClinVar RCV002420173, Uncertain significance, Inborn genetic diseases
- Q75H (p.Gln75His), NCI-TCGA Cosmic COSV6171, REVEL 0.43, CADD 20.30, Variant assessed as somatic; moderate impact.
- N76S (p.Asn76Ser), rs2520900734, ClinGen CA414527203, ClinVar RCV002820802, Uncertain significance, Mucopolysaccharidosis, MPS-II
- A77D (p.Ala77Asp), rs2520900702, ClinGen CA414527184, ClinVar RCV003066396, Pathogenic, Mucopolysaccharidosis, MPS-II
- A79E (p.Ala79Glu), UniProt VAR 007318, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- A79G (p.Ala79Gly), rs368513342, ClinGen CA10537720, ClinVar RCV001514532, ClinVar RCV004037927, REVEL 0.87, CADD 24.70, Benign/Likely benign, Mucopolysaccharidosis, MPS-II; Inborn genetic diseases
- A79V (p.Ala79Val), rs368513342, ClinGen CA10537721, ClinVar RCV001825437, ClinVar RCV002313580, REVEL 0.69, CADD 20.20, Uncertain significance, Mucopolysaccharidosis, MPS-II; Inborn genetic diseases
- Q80* (p.Gln80Ter), Ensembl rs1569560527, Pathogenic
- Q80R (p.Gln80Arg), rs2520900502, ClinGen CA414527123, ClinVar RCV002430660, ClinVar RCV003098851, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II; Inborn genetic diseases
- Q81* (p.Gln81Ter), rs2520897240, ClinGen CA414527009, ClinVar RCV003140688, Pathogenic
- A82E (p.Ala82Glu), UniProt VAR 008999, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- A82T (p.Ala82Thr), rs2520897215, ClinGen CA414526988, ClinVar RCV004526464, Uncertain significance, not specified
- A82V (p.Ala82Val), UniProt VAR 026918, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- V83G (p.Val83Gly), rs1569560525, ClinGen CA414526958, ClinVar RCV002535424, ClinVar RCV005251181, AlphaMissense 0.85, MetaLR 1.00, Conflicting interpretations, Mucopolysaccharidosis, MPS-II; not provided
- C84* (p.Cys84Ter), rs1557340286, ClinGen CA414526935, ClinVar RCV000593133, ClinVar RCV004596301, AlphaMissense 1.00, MetaLR 1.00, Pathogenic
- C84W (p.Cys84Trp), rs1557340286, ClinGen CA414526933, ClinVar RCV001291744, TOPMed rs1557340286, AlphaMissense 1.00, MetaLR 1.00, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- A85S (p.Ala85Ser), UniProt VAR 026919, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- A85T (p.Ala85Thr), rs113993949, ClinGen CA331781, NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, AlphaMissense 0.71, MetaLR 0.93, Pathogenic/Likely pathogenic, not provided; Mucopolysaccharidosis, MPS-II
- P86L (p.Pro86Leu), rs1557340280, ClinGen CA414526900, ClinVar RCV000632180, ClinVar RCV002458004, AlphaMissense 0.91, MetaLR 1.00, Pathogenic, not provided; Mucopolysaccharidosis, MPS-II; Mucopolysaccharidosis, MPS-III-A
- P86Q (p.Pro86Gln), UniProt VAR 007321, Pathogenic, Mucopolysaccharidosis, MPS-II
- P86R (p.Pro86Arg), rs1557340280, ClinGen CA414526902, ClinVar RCV001291743, UniProt VAR 007322, REVEL 0.99, AlphaMissense 0.91, Pathogenic, Mucopolysaccharidosis, MPS-II
- S87N (p.Ser87Asn), UniProt VAR 007323, Conflicting interpretations, Mucopolysaccharidosis, MPS-II
- R88C (p.Arg88Cys), rs398123249, ClinGen CA220494, ClinVar RCV000177014, ClinVar RCV000790676, AlphaMissense 0.95, MetaLR 1.00, Pathogenic, not provided; Mucopolysaccharidosis, MPS-II
- R88G (p.Arg88Gly), UniProt VAR 026920, Pathogenic, Mucopolysaccharidosis, MPS-II
- R88H (p.Arg88His), rs2089497431, ClinGen CA414526862, ClinVar RCV001222779, UniProt VAR 007325, AlphaMissense 0.94, MetaLR 1.00, Pathogenic/Likely pathogenic, Mucopolysaccharidosis, MPS-II
- R88L (p.Arg88Leu), UniProt VAR 007326, Pathogenic, Mucopolysaccharidosis, MPS-II
- R88P (p.Arg88Pro), UniProt VAR 007327, Pathogenic, Mucopolysaccharidosis, MPS-II
- V89F (p.Val89Phe), UniProt VAR 026921, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- V89G (p.Val89Gly), rs2520896995, ClinGen CA414526825, ClinVar RCV002437287, Uncertain significance, Inborn genetic diseases
- V89I (p.Val89Ile), rs1557340275, NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, TOPMed rs1557340275, REVEL 0.49, CADD 16.90, Uncertain significance, Mucopolysaccharidosis, MPS-II
- S90C (p.Ser90Cys), rs2520896970, ClinGen CA414526810, ClinVar RCV002428983, Uncertain significance, Inborn genetic diseases
- F91L (p.Phe91Leu), rs2520896951, ClinGen CA414526778, ClinVar RCV002707255, Uncertain significance, Inborn genetic diseases
- L92P (p.Leu92Pro), rs2089497300, ClinGen CA414526758, ClinVar RCV001291036, UniProt VAR 007328, AlphaMissense 0.99, MetaLR 0.99, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- G94D (p.Gly94Asp), UniProt VAR 007329, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- R95G (p.Arg95Gly), UniProt VAR 026922, Pathogenic/Likely pathogenic, not provided; Mucopolysaccharidosis, MPS-II
- R95T (p.Arg95Thr), UniProt VAR 026923, Pathogenic, Mucopolysaccharidosis, MPS-II
- R95W (p.Arg95Trp), rs2089497268, ClinGen CA414526688, ClinVar RCV001290995, Ensembl rs2089497268, AlphaMissense 0.74, MetaLR 0.98, Pathogenic, Mucopolysaccharidosis, MPS-II
- R96G (p.Arg96Gly), Ensembl rs2089497193, REVEL 0.93, CADD 25.30, Uncertain significance, not provided
- P97A (p.Pro97Ala), gnomAD rs1557340273, Uncertain significance, Mucopolysaccharidosis, MPS-III-A
- P97T (p.Pro97Thr), rs1557340273, ClinGen CA414526622, ClinVar RCV001887738, ClinVar RCV003375375, REVEL 0.95, CADD 26.10, Uncertain significance, not provided; Mucopolysaccharidosis, MPS-II; Inborn genetic diseases
- D98A (p.Asp98Ala), TOPMed rs2089497099
- D98G (p.Asp98Gly), TOPMed rs2089497099, REVEL 0.91, CADD 28.00
- T99I (p.Thr99Ile), TOPMed rs2089497015, REVEL 0.95, CADD 26.20
- T100I (p.Thr100Ile), TOPMed rs2089496924, gnomAD rs2089496924, REVEL 0.87, CADD 24.00
- T100P (p.Thr100Pro), ExAC rs782118903, gnomAD rs782118903, REVEL 0.92, CADD 25.00
- R101C (p.Arg101Cys), rs782738754, ClinGen CA10537707, ClinVar RCV000353621, ClinVar RCV001088215, REVEL 0.93, CADD 28.00, Conflicting interpretations, not provided; Mucopolysaccharidosis, MPS-II
- R101H (p.Arg101His), rs1391120386, ClinGen CA414526526, NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, REVEL 0.72, CADD 20.50, Uncertain significance, not provided; Inborn genetic diseases
- R101L (p.Arg101Leu), 1000Genomes rs1391120386, TOPMed rs1391120386, gnomAD rs1391120386, Uncertain significance
- L102P (p.Leu102Pro), rs1557340261, ClinGen CA414526516, ClinVar RCV001837738, gnomAD rs1557340261, AlphaMissense 0.82, MetaLR 0.96, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- L102Q (p.Leu102Gln), gnomAD rs1557340261, REVEL 0.96, AlphaMissense 0.82, Uncertain significance, not provided
- L102R (p.Leu102Arg), UniProt VAR 007330, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- Y103* (p.Tyr103Ter), rs1174495581, ClinGen CA414526483, ClinVar RCV003126330, ClinVar RCV004596571, Pathogenic
- Y103D (p.Tyr103Asp), rs2089496667, ClinGen CA414526498, ClinVar RCV001290998, Ensembl rs2089496667, AlphaMissense 0.95, MetaLR 0.97, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- D104E (p.Asp104Glu), Ensembl rs2124063377, Likely benign
- D104N (p.Asp104Asn), rs1557340258, gnomAD rs1557340258, REVEL 0.70, CADD 24.40, Uncertain significance, not specified; Mucopolysaccharidosis, MPS-II
- F105L (p.Phe105Leu), rs2124063363, ClinGen CA414526426, ClinVar RCV002704156, Ensembl rs2124063363, AlphaMissense 0.95, MetaLR 0.98, Uncertain significance, Inborn genetic diseases
- N106K (p.Asn106Lys), rs2089496498, ClinGen CA414526396, ClinVar RCV002714309, Uncertain significance, Inborn genetic diseases
- S107C (p.Ser107Cys), ExAC rs782067898, gnomAD rs782067898
- Y108* (p.Tyr108Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact., in MPS2
- Y108C (p.Tyr108Cys), UniProt VAR 007331, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- Y108D (p.Tyr108Asp), rs2520896190, ClinGen CA414526359, ClinVar RCV002289443, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- Y108H (p.Tyr108His), rs2520896190, ClinGen CA414526363, ClinVar RCV003238948, Uncertain significance, not provided
- Y108S (p.Tyr108Ser), UniProt VAR 026924, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- W109* (p.Trp109Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- R110G (p.Arg110Gly), rs2124063287, ClinGen CA414526288, ClinVar RCV001378371, ClinVar RCV004720886, AlphaMissense 0.97, MetaLR 0.95, Pathogenic/Likely pathogenic, not provided; Mucopolysaccharidosis, MPS-II
- V111A (p.Val111Ala), Ensembl rs2124063265
- V111L (p.Val111Leu), rs1602748386, ClinGen CA414526253, ClinVar RCV000795807, Ensembl rs1602748386, AlphaMissense 0.11, MetaLR 0.84, Uncertain significance, Mucopolysaccharidosis, MPS-II
- H112L (p.His112Leu), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10055, Variant assessed as somatic; moderate impact.
- A113S (p.Ala113Ser), NCI-TCGA Cosmic COSV6171, Ensembl rs2124063209, Uncertain significance
- A113T (p.Ala113Thr), rs2124063209, ClinGen CA414526199, NCI-TCGA Cosmic COSV6171, cosmic curated COSV61713, REVEL 0.40, CADD 16.90, Uncertain significance, Mucopolysaccharidosis, MPS-II
- N115Y (p.Asn115Tyr), UniProt VAR 007332, Pathogenic, Mucopolysaccharidosis, MPS-II
- F116V (p.Phe116Val), rs2124063192, ClinGen CA414526142, ClinVar RCV002027870, Ensembl rs2124063192, AlphaMissense 0.58, MetaLR 0.90, Uncertain significance, Mucopolysaccharidosis, MPS-II
- S117F (p.Ser117Phe), rs2520895937, ClinGen CA414526109, ClinVar RCV003324317, REVEL 0.84, CADD 24.60, Uncertain significance, not specified
- S117Y (p.Ser117Tyr), UniProt VAR 026926, Likely pathogenic, Mucopolysaccharidosis, MPS-II
- T118I (p.Thr118Ile), rs2520895871, ClinGen CA414526087, ClinVar RCV003146149, ClinVar RCV003420582, Pathogenic/Likely pathogenic, IDS-related disorder; Mucopolysaccharidosis, MPS-II
- T118S (p.Thr118Ser), rs2089496220, ClinGen CA414526091, ClinVar RCV001923583, ClinVar RCV004616878, REVEL 0.85, CADD 23.70, Uncertain significance, Mucopolysaccharidosis, MPS-II; Inborn genetic diseases
- P120H (p.Pro120His), rs193302911, ClinGen CA349872, ClinVar RCV000205759, UniProt VAR 007334, AlphaMissense 0.88, MetaLR 1.00, Pathogenic, in MPS2
Public IDS analysis runs
- IDS analysis run — IDS (897 variants) — completed 2026-08-19