LDB3 (LIM domain-binding protein 3) variants and mutations
LDB3 (also known as LIM domain-binding protein 3) is a human protein-coding gene encoding a LIM domain-binding protein 3 protein. It organizes Z-disc protein complexes and helps maintain sarcomere integrity during repeated muscle contraction. Pathogenic variants can cause myofibrillar myopathy and dilated or other forms of cardiomyopathy. This analysis covers 1,449 LDB3 variants and mutations. Of these, 77% have computational variant effect predictions. Disease context includes myofibrillar myopathy 4, hypertrophic cardiomyopathy, and Late-onset distal myopathy, Markesbery-Griggs type. Example LDB3 variants include S2P, S2T, and S2Y.
Variant analysis overview
- Gene: LDB3
- Protein: LIM domain-binding protein 3
- UniProt accession: O75112
- Organism: Homo sapiens
- Variants analyzed: 1449
- Variant scope: all variants
- Completed: 2026-08-20
Variant and mutation evidence
- Variant composition: 1,207 unspecified-consequence records; 11 natural variant; 92 missense variants; 114 synonymous variants; 2 stop-gained variants; 1 in-frame insertions; 10 frameshift variants; 3 splice-region variants; 7 in-frame deletions; 2 substitution
- Prediction scores: 1,119 variants have prediction scores (77% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: myofibrillar myopathy 4, hypertrophic cardiomyopathy, Late-onset distal myopathy, Markesbery-Griggs type, left ventricular noncompaction, cardiomyopathy, dilated, 2l, atrial fibrillation, dilated cardiomyopathy, Rare familial disorder with hypertrophic cardiomyopathy, familial isolated dilated cardiomyopathy, myofibrillar myopathy, Abnormality of the cardiovascular system, cardiomyopathy.
Protein structure and variant hotspots
- Protein features: 4 domains; 8 post-translational modification sites.
- Structural context: 490 variants have structural context.
- PTM context: 24 variants overlap post-translational modification sites.
- Experimental data: 83 protein positions have experimental scores. Source: LDB3 PDZ domain domainome 1.0.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable LDB3 variants
Examples include S2P, S2T, S2Y, S2F, Y3Y, S4N, S4R, S4T. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- S2P (p.Ser2Pro), TOPMed rs1564626023, REVEL 0.11, AlphaMissense 0.16, Uncertain significance, Cardiovascular phenotype
- S2T (p.Ser2Thr), rs1564626023, ClinGen CA377448663, ClinVar RCV000687165, TOPMed rs1564626023, AlphaMissense 0.16, MetaLR 0.09, Uncertain significance, Myofibrillar myopathy 4
- S2Y (p.Ser2Tyr), rs1564626030, ClinGen CA377448667, ClinVar RCV000770134, Ensembl rs1564626030, REVEL 0.35, CADD 26.70, Uncertain significance, Cardiomyopathy
- S2F (p.Ser2Phe), gnomAD 10-86668696-C-T, REVEL 0.28, CADD 27.50
- Y3Y (p.Tyr3Tyr), gnomAD 10-86668700-C-T, CADD 13.20
- S4N (p.Ser4Asn), rs766405051, ClinGen CA5584560, ClinVar RCV001536972, ClinVar RCV001873806, REVEL 0.03, CADD 22.80, Conflicting interpretations, Cardiovascular phenotype; not provided; Myofibrillar myopathy 4
- S4R (p.Ser4Arg), rs727505295, ClinGen CA185660, ClinVar RCV000156828, ClinVar RCV003611499, REVEL 0.32, CADD 29.40, Uncertain significance, not specified; Myofibrillar myopathy 4
- S4T (p.Ser4Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S4I (p.Ser4Ile), gnomAD 10-86668702-G-T, REVEL 0.22, CADD 28.30
- V5M (p.Val5Met), rs773170985, ClinGen CA5584562, ClinVar RCV001774003, ClinVar RCV002034481, REVEL 0.59, CADD 31.00, Uncertain significance, Myofibrillar myopathy 4; Dilated cardiomyopathy 1C; Cardiovascular phenotype
- V5V (p.Val5Val), gnomAD 10-86668706-G-A, CADD 13.50
- T6I (p.Thr6Ile), gnomAD 10-86668708-C-T, REVEL 0.20, CADD 25.90
- L7L (p.Leu7Leu), gnomAD 10-86668710-C-T, CADD 13.60
- L7P (p.Leu7Pro), gnomAD 10-86668711-T-C, REVEL 0.67, CADD 32.00
- T8N (p.Thr8Asn), rs1060501317, ClinGen CA16613180, ClinVar RCV000462573, ClinVar RCV000786156, REVEL 0.04, CADD 17.90, Uncertain significance, Myofibrillar myopathy 4; not provided
- T8P (p.Thr8Pro), cosmic curated COSV10502, REVEL 0.03, CADD 20.90
- T8S (p.Thr8Ser), gnomAD 10-86668713-A-T, REVEL 0.04, CADD 18.90
- T8T (p.Thr8Thr), rs1269874524, gnomAD 10-86668715-T-G, CADD 4.98
- G9R (p.Gly9Arg), NCI-TCGA Cosmic COSV9955, cosmic curated COSV99555, REVEL 0.58, CADD 32.00, Variant assessed as somatic; moderate impact.
- G9V (p.Gly9Val), rs2492473660, ClinGen CA377448709, ClinVar RCV002428994, NCI-TCGA Cosmic COSV5394, Uncertain significance, Cardiovascular phenotype
- G9G (p.Gly9Gly), rs547733235, gnomAD 10-86668718-G-C, CADD 13.50
- P10H (p.Pro10His), NCI-TCGA Cosmic COSV9955, cosmic curated COSV99554, Variant assessed as somatic; moderate impact.
- P10A (p.Pro10Ala), gnomAD 10-86668719-C-G, REVEL 0.36, CADD 26.20
- P10S (p.Pro10Ser), gnomAD 10-86668719-C-T, REVEL 0.41, CADD 27.10
- P10R (p.Pro10Arg), gnomAD 10-86668720-C-G, REVEL 0.46, CADD 28.90
- P10P (p.Pro10Pro), rs766817285, gnomAD 10-86668721-C-G, CADD 7.92
- G11R (p.Gly11Arg), rs370493508, ClinGen CA5584565, ClinVar RCV001305116, ESP rs370493508, REVEL 0.43, CADD 32.00, Uncertain significance, Myofibrillar myopathy 4
- G11W (p.Gly11Trp), rs370493508, ClinGen CA377448717, ClinVar RCV003612486, REVEL 0.47, CADD 32.00, Uncertain significance, Myofibrillar myopathy 4
- G11E (p.Gly11Glu), gnomAD 10-86668723-G-A, REVEL 0.26, CADD 28.00
- G11G (p.Gly11Gly), rs1489243724, gnomAD 10-86668724-G-A, CADD 10.80
- P12H (p.Pro12His), cosmic curated COSV53948
- P12L (p.Pro12Leu), rs2492473876, ClinGen CA377448723, ClinVar RCV004517255, cosmic curated COSV53939, REVEL 0.54, CADD 29.50, Uncertain significance, Cardiovascular phenotype
- P12S (p.Pro12Ser), Ensembl rs113065084, REVEL 0.51, CADD 27.90
- P12T (p.Pro12Thr), gnomAD 10-86668725-C-A, REVEL 0.55, CADD 26.80
- P12P (p.Pro12Pro), rs1564626136, gnomAD 10-86668727-C-A, CADD 14.30
- W13C (p.Trp13Cys), gnomAD rs1844289659, REVEL 0.58, CADD 33.00
- W13* (p.Trp13Ter), gnomAD 10-86668729-G-A, CADD 44.00
- G14G (p.Gly14Gly), rs563734579, gnomAD 10-86668733-C-T, CADD 14.30
- F15L (p.Phe15Leu), ExAC rs760017084, gnomAD rs760017084, REVEL 0.69, CADD 32.00
- R16C (p.Arg16Cys), rs1844290057, ClinGen CA377448750, cosmic curated COSV53944, ClinVar RCV002895061, REVEL 0.47, CADD 32.00, Uncertain significance, Myofibrillar myopathy 4
- R16H (p.Arg16His), rs767986134, ClinGen CA5584567, ClinVar RCV001244847, ClinVar RCV002327594, REVEL 0.57, CADD 32.00, Uncertain significance, Cardiovascular phenotype; Myofibrillar myopathy 4
- L17P (p.Leu17Pro), rs2132320405, ClinGen CA377448756, ClinVar RCV002026668, Ensembl rs2132320405, AlphaMissense 1.00, MetaLR 0.35, Uncertain significance, Myofibrillar myopathy 4
- L17M (p.Leu17Met), gnomAD 10-86668740-C-A, REVEL 0.34, CADD 24.30
- L17L (p.Leu17Leu), gnomAD 10-86668742-G-T, CADD 9.38
- p.Leu17 Gln18insPro, gnomAD 10-86668742-G-GCC, CADD 21.80
- Q18H (p.Gln18His), rs149348427, ClinGen CA308654, ClinVar RCV000183544, ClinVar RCV000763672, REVEL 0.31, CADD 24.20, Conflicting interpretations, Cardiovascular phenotype; Dilated cardiomyopathy 1C; Myofibrillar myopathy 4
- Q18P (p.Gln18Pro), TOPMed rs1844290505
- Q18Q (p.Gln18Gln), rs149348427, gnomAD 10-86668745-G-A, CADD 10.50
- G19A (p.Gly19Ala), rs753314972, ClinGen CA5584570, ClinVar RCV001767037, ClinVar RCV002032843, REVEL 0.54, AlphaMissense 1.00, Uncertain significance, Cardiovascular phenotype; not provided; Myofibrillar myopathy 4
- G19E (p.Gly19Glu), rs753314972, ClinGen CA377448767, ClinVar RCV001205109, ExAC rs753314972, AlphaMissense 1.00, MetaLR 0.34, Uncertain significance, Myofibrillar myopathy 4
- G19R (p.Gly19Arg), rs777413488, ClinGen CA5584569, ClinVar RCV001242293, ClinVar RCV002348825, REVEL 0.54, CADD 32.00, Uncertain significance, Cardiovascular phenotype; Dilated cardiomyopathy 1C; Myofibrillar myopathy 4
- G19W (p.Gly19Trp), rs777413488, ClinGen CA377448765, ClinVar RCV000795954, ClinVar RCV004639356, REVEL 0.56, CADD 32.00, Uncertain significance, Cardiovascular phenotype; Myofibrillar myopathy 4
- G19G (p.Gly19Gly), rs756773220, gnomAD 10-86668748-G-A, CADD 8.47
- G20D (p.Gly20Asp), rs1844291597, ClinGen CA377448772, ClinVar RCV001923875, TOPMed rs1844291597, REVEL 0.65, CADD 31.00, Uncertain significance, Myofibrillar myopathy 4
- G20S (p.Gly20Ser), rs2492474388, ClinGen CA377448769, ClinVar RCV003613287, REVEL 0.59, CADD 32.00, Uncertain significance, Myofibrillar myopathy 4
- G20A (p.Gly20Ala), rs1308589918, gnomAD 10-86668744-AG-A, CADD 25.10
- G20K (p.Gly20Lys), gnomAD 10-86668746-G-GGC, CADD 32.00
- G20G (p.Gly20Gly), gnomAD 10-86668751-C-T, CADD 17.90
- K21Q (p.Lys21Gln), NCI-TCGA Cosmic COSV5394, Variant assessed as somatic; high impact.
- K21K (p.Lys21Lys), rs1165515256, gnomAD 10-86668754-G-A, CADD 13.00
- D22E (p.Asp22Glu), rs1261515174, ClinGen CA377448789, ClinVar RCV000853154, ClinVar RCV003424373, REVEL 0.35, CADD 26.10, Uncertain significance, not provided; Primary familial hypertrophic cardiomyopathy
- D22G (p.Asp22Gly), gnomAD 10-86668745-G-GGG, CADD 33.00
- F23S (p.Phe23Ser), gnomAD 10-86668759-T-C, REVEL 0.55, CADD 32.00
- N24I (p.Asn24Ile), gnomAD rs1351889251, REVEL 0.54, CADD 29.60, Uncertain significance, Myofibrillar myopathy 4
- N24K (p.Asn24Lys), rs1323002546, ClinGen CA377448805, ClinVar RCV000687898, ClinVar RCV001091334, REVEL 0.29, CADD 24.30, Uncertain significance, Cardiovascular phenotype; not provided; Myofibrillar myopathy 4
- N24N (p.Asn24Asn), gnomAD 10-86668763-C-T, CADD 11.70
- M25I (p.Met25Ile), Ensembl rs1844292439
- M25T (p.Met25Thr), rs1422946564, ClinGen CA377448812, ClinVar RCV003047679, ClinVar RCV005869984, REVEL 0.49, CADD 29.60, Uncertain significance, not provided; Myofibrillar myopathy 4
- M25V (p.Met25Val), gnomAD 10-86668764-A-G, REVEL 0.31, CADD 26.90
- P26S (p.Pro26Ser), rs778865072, ClinGen CA5584572, ClinVar RCV001768464, ClinVar RCV002540245, REVEL 0.48, CADD 27.20, Uncertain significance, not provided; Myofibrillar myopathy 4
- P26L (p.Pro26Leu), gnomAD 10-86668768-C-T, REVEL 0.48, CADD 30.00
- L27F (p.Leu27Phe), rs1554844343, ClinGen CA377448823, ClinVar RCV000521458, Ensembl rs1554844343, REVEL 0.36, CADD 27.00, Uncertain significance, not provided
- L27P (p.Leu27Pro), rs1057517864, ClinGen CA16042803, ClinVar RCV000414048, ClinVar RCV000800067, REVEL 0.68, CADD 32.00, Uncertain significance, Cardiovascular phenotype; not specified; Myofibrillar myopathy 4
- L27V (p.Leu27Val), gnomAD 10-86668770-C-G, REVEL 0.26, CADD 25.90
- L27L (p.Leu27Leu), rs1554844351, gnomAD 10-86668772-C-G, CADD 12.80
- T28S (p.Thr28Ser), Ensembl rs1844293701, REVEL 0.28, CADD 26.40, Uncertain significance, Myofibrillar myopathy 4
- I29L (p.Ile29Leu), gnomAD 10-86668776-A-C, REVEL 0.37, CADD 29.70
- I29V (p.Ile29Val), gnomAD 10-86668776-A-G, REVEL 0.12, CADD 27.30
- I29I (p.Ile29Ile), gnomAD 10-86668778-C-T, CADD 12.70
- S30C (p.Ser30Cys), rs1844293917, ClinGen CA377448843, ClinVar RCV002811412, AlphaMissense 0.99, MetaLR 0.33, Uncertain significance, Myofibrillar myopathy 4
- S30Y (p.Ser30Tyr), rs1844293917, ClinGen CA377448842, ClinVar RCV001202464, Ensembl rs1844293917, AlphaMissense 0.99, MetaLR 0.33, Uncertain significance, Myofibrillar myopathy 4
- R31G (p.Arg31Gly), rs367792378, ClinGen CA377448845, ClinVar RCV001347909, ClinVar RCV004629591, REVEL 0.40, CADD 27.60, Uncertain significance, Cardiovascular phenotype; not specified; Myofibrillar myopathy 4
- R31L (p.Arg31Leu), TOPMed rs1410128172, gnomAD rs1410128172, Uncertain significance
- R31Q (p.Arg31Gln), rs1410128172, ClinGen CA377448846, NCI-TCGA Cosmic COSV5395, cosmic curated COSV53951, REVEL 0.32, CADD 34.00, Uncertain significance, Myofibrillar myopathy 4
- R31W (p.Arg31Trp), rs367792378, ClinGen CA308659, ClinVar RCV000183545, ClinVar RCV000469897, REVEL 0.41, CADD 32.00, Uncertain significance, Cardiovascular phenotype; not specified; not provided
- R31R (p.Arg31Arg), rs1564626245, gnomAD 10-86668784-G-A, CADD 24.10
- I32V (p.Ile32Val), rs2492563077, ClinGen CA377450980, ClinVar RCV003503342, Uncertain significance, Myofibrillar myopathy 4
- T33I (p.Thr33Ile), cosmic curated COSV99554, Ensembl rs1844982244, REVEL 0.35, CADD 26.10
- T33S (p.Thr33Ser), ExAC rs777894465, gnomAD rs777894465, REVEL 0.11, CADD 23.80
- P34Q (p.Pro34Gln), cosmic curated COSV99555
- P34R (p.Pro34Arg), rs2492563180, ClinGen CA377451019, ClinVar RCV003504038, REVEL 0.54, CADD 25.70, Uncertain significance, Myofibrillar myopathy 4
- P34T (p.Pro34Thr), TOPMed rs1844982695
- G35D (p.Gly35Asp), Ensembl rs1844983187, REVEL 0.69, CADD 29.40
- G35S (p.Gly35Ser), NCI-TCGA Cosmic COSV5394, cosmic curated COSV53940, Variant assessed as somatic; moderate impact.
- G35G (p.Gly35Gly), gnomAD 10-86679378-C-G, CADD 8.85
- S36R (p.Ser36Arg), rs2132360019, NCI-TCGA TCGA novel, ClinGen CA377451058, ClinVar RCV001891401, AlphaMissense 1.00, MetaLR 0.47, Uncertain significance, Myofibrillar myopathy 4
- S36N (p.Ser36Asn), gnomAD 10-86679380-G-A, REVEL 0.46, CADD 28.30
- K37M (p.Lys37Met), rs2132360031, ClinGen CA377451067, ClinVar RCV001882961, Ensembl rs2132360031, AlphaMissense 0.95, MetaLR 0.29, Uncertain significance, Myofibrillar myopathy 4
- K37R (p.Lys37Arg), rs2132360031, ClinGen CA377451066, ClinVar RCV003503545, AlphaMissense 0.95, MetaLR 0.29, Uncertain significance, Myofibrillar myopathy 4
- A38T (p.Ala38Thr), ExAC rs771189193, gnomAD rs771189193, REVEL 0.77, CADD 31.00
- A38A (p.Ala38Ala), rs556222085, gnomAD 10-86679387-A-C, CADD 2.19
- A39P (p.Ala39Pro), rs1844983837, ClinGen CA377451087, ClinVar RCV001232957, Ensembl rs1844983837, AlphaMissense 0.99, MetaLR 0.49, Uncertain significance, Myofibrillar myopathy 4
- A39T (p.Ala39Thr), gnomAD 10-86679388-G-A, REVEL 0.40, CADD 28.60
- A39A (p.Ala39Ala), rs2132360061, gnomAD 10-86679390-C-G, CADD 8.75
- Q40* (p.Gln40Ter), cosmic curated COSV53946
- Q40H (p.Gln40His), Ensembl rs2132360072
- S41S (p.Ser41Ser), rs147548646, gnomAD 10-86679396-C-T, CADD 8.27
- Q42E (p.Gln42Glu), Ensembl rs2132360100
- Q42H (p.Gln42His), TOPMed rs1177908121, gnomAD rs1177908121, REVEL 0.10, CADD 23.70
- Q42P (p.Gln42Pro), 1000Genomes rs2132360110, REVEL 0.18, CADD 25.70
- Q42S (p.Gln42Ser), gnomAD 10-86679394-TCCCA, CADD 32.00
- L43F (p.Leu43Phe), cosmic curated COSV53947, REVEL 0.43, CADD 23.60
- L43V (p.Leu43Val), gnomAD 10-86679400-C-G, REVEL 0.17, CADD 16.00
- L43L (p.Leu43Leu), rs772734712, gnomAD 10-86679402-C-T, CADD 9.29
- S44R (p.Ser44Arg), gnomAD 10-86679405-C-G, REVEL 0.06, CADD 22.80
- S44S (p.Ser44Ser), gnomAD 10-86679405-C-T, CADD 11.40
- Q45* (p.Gln45Ter), rs1057524744, ClinGen CA16605696, ClinVar RCV000422854, Ensembl rs1057524744, Uncertain significance
- G46C (p.Gly46Cys), ExAC rs776046497, TOPMed rs776046497, gnomAD rs776046497, REVEL 0.58, CADD 31.00, Uncertain significance, Myofibrillar myopathy 4; Cardiovascular phenotype
- G46R (p.Gly46Arg), gnomAD 10-86679409-G-C, REVEL 0.64, CADD 29.20
- G46D (p.Gly46Asp), gnomAD 10-86679410-G-A, REVEL 0.64, CADD 28.10
- G46V (p.Gly46Val), gnomAD 10-86679410-G-T, REVEL 0.60, CADD 27.90
- G46G (p.Gly46Gly), gnomAD 10-86679411-T-G, CADD 3.68
- D47E (p.Asp47Glu), TOPMed rs1331679700
- D47N (p.Asp47Asn), rs397517212, ClinGen CA136503, ClinVar RCV000038725, ClinVar RCV000811533, REVEL 0.73, CADD 31.00, Uncertain significance, Cardiovascular phenotype; not specified; not provided
- L48F (p.Leu48Phe), gnomAD 10-86679415-C-T, REVEL 0.07, CADD 19.80
- L48R (p.Leu48Arg), gnomAD 10-86679416-T-G, REVEL 0.42, CADD 27.30
- L48L (p.Leu48Leu), rs397517213, gnomAD 10-86679417-C-A, CADD 0.63
- V49L (p.Val49Leu), rs200645175, ClinGen CA5584602, ClinVar RCV001071537, ClinVar RCV002480445, REVEL 0.36, CADD 25.80, Uncertain significance, not specified; Myofibrillar myopathy 4; Cardiovascular phenotype
- V49M (p.Val49Met), rs200645175, ClinGen CA5584603, ClinVar RCV001326988, ClinVar RCV002070150, REVEL 0.36, CADD 26.70, Uncertain significance, Cardiovascular phenotype; Myofibrillar myopathy 4; not provided
- V49V (p.Val49Val), rs45591834, gnomAD 10-86679420-G-C, CADD 9.33
- V50A (p.Val50Ala), rs1844986603, ClinGen CA377451229, ClinVar RCV001306227, Ensembl rs1844986603, AlphaMissense 0.66, MetaLR 0.20, Uncertain significance, Myofibrillar myopathy 4
- A51V (p.Ala51Val), rs1408157154, ClinGen CA377451242, ClinVar RCV002630908, TOPMed rs1408157154, AlphaMissense 0.76, MetaLR 0.29, Uncertain significance, Myofibrillar myopathy 4
- A51A (p.Ala51Ala), rs1161225357, gnomAD 10-86679426-C-T, CADD 11.80
- I52T (p.Ile52Thr), rs1449865053, ClinGen CA377451247, ClinVar RCV001946108, ClinVar RCV002397952, REVEL 0.60, CADD 27.30, Uncertain significance, Dilated cardiomyopathy 1C; Myofibrillar myopathy 4; Cardiovascular phenotype
- D53G (p.Asp53Gly), rs935307586, ClinGen CA211209322, ClinVar RCV002041303, ClinVar RCV004641895, REVEL 0.70, CADD 25.50, Uncertain significance, Myofibrillar myopathy 4; Cardiovascular phenotype
- D53N (p.Asp53Asn), rs2132360328, ClinGen CA377451254, ClinVar RCV001768447, ClinVar RCV001882855, REVEL 0.32, CADD 26.00, Uncertain significance, not provided; Myofibrillar myopathy 4
- D53D (p.Asp53Asp), rs200114285, gnomAD 10-86679432-C-T, CADD 2.05
- G54R (p.Gly54Arg), rs201786090, ClinGen CA377451271, ClinVar RCV001963459, 1000Genomes rs201786090, AlphaMissense 0.48, MetaLR 0.39, Uncertain significance, Myofibrillar myopathy 4
- G54S (p.Gly54Ser), rs201786090, ClinGen CA221472, ClinVar RCV000079441, ClinVar RCV000706758, REVEL 0.50, AlphaMissense 0.48, Uncertain significance, Cardiovascular phenotype; not provided; Myofibrillar myopathy 4
- G54D (p.Gly54Asp), gnomAD 10-86679434-G-A, REVEL 0.57, CADD 27.90
- G54G (p.Gly54Gly), rs757856121, gnomAD 10-86679435-C-T, CADD 6.64
- V55A (p.Val55Ala), gnomAD rs1339140048, Uncertain significance, Cardiovascular phenotype
- V55I (p.Val55Ile), rs3740343, ClinGen CA136549, cosmic curated COSV53952, ClinVar RCV000038739, REVEL 0.04, CADD 19.60, Benign/Likely benign, Cardiovascular phenotype; Dilated cardiomyopathy 1C; Myofibrillar myopathy 4
- V55V (p.Val55Val), rs1222411686, gnomAD 10-86679438-C-A, CADD 9.57
- N56S (p.Asn56Ser), rs751482077, ClinGen CA5584605, ClinVar RCV001214500, ClinVar RCV004726972, REVEL 0.09, CADD 18.10, Uncertain significance, not provided; Cardiovascular phenotype; Myofibrillar myopathy 4
- T57T (p.Thr57Thr), rs754796151, gnomAD 10-86679444-A-G, CADD 7.86
- D58N (p.Asp58Asn), rs730880127, ClinGen CA346419, ClinVar RCV000157286, ClinVar RCV001337557, REVEL 0.23, CADD 28.80, Uncertain significance, Cardiovascular phenotype; Myofibrillar myopathy 4
- D58D (p.Asp58Asp), rs781026398, gnomAD 10-86679447-C-T, CADD 6.06
- T59A (p.Thr59Ala), rs1219221888, ClinGen CA377451323, ClinVar RCV003846448, ClinVar RCV005662751, REVEL 0.07, CADD 21.90, Conflicting interpretations, Myofibrillar myopathy 4; Cardiovascular phenotype
- T59I (p.Thr59Ile), gnomAD 10-86679449-C-T, REVEL 0.25, CADD 23.80
- M60L (p.Met60Leu), rs747835472, ExAC rs747835472, gnomAD rs747835472, REVEL 0.34, CADD 26.70, Uncertain significance, Myofibrillar myopathy 4
- T61I (p.Thr61Ile), rs2492564614, ClinGen CA377451354, ClinVar RCV003337993, REVEL 0.56, CADD 25.90, Uncertain significance, Myofibrillar myopathy 4
- T61P (p.Thr61Pro), ExAC rs757553784, gnomAD rs757553784, REVEL 0.57, CADD 28.60
- T61T (p.Thr61Thr), rs1466464578, gnomAD 10-86679456-C-A, CADD 9.54
- H62Y (p.His62Tyr), rs779234633, ClinGen CA5584610, ClinVar RCV000494440, ClinVar RCV003766776, REVEL 0.59, CADD 25.60, Uncertain significance, not provided; Myofibrillar myopathy 4
- L63P (p.Leu63Pro), cosmic curated COSV10454, REVEL 0.58, CADD 31.00
- E64K (p.Glu64Lys), NCI-TCGA Cosmic COSV5394, cosmic curated COSV53949, TOPMed rs1844991080, REVEL 0.54, CADD 32.00, Variant assessed as somatic; moderate impact.
- A65T (p.Ala65Thr), Ensembl rs1589618018, REVEL 0.51, CADD 29.50
- A65A (p.Ala65Ala), gnomAD 10-86679468-C-A, CADD 9.95
- Q66* (p.Gln66Ter), rs1554849100, ClinGen CA377451403, ClinVar RCV000639874, Ensembl rs1554849100, Pathogenic
- Q66R (p.Gln66Arg), cosmic curated COSV53950
- N67S (p.Asn67Ser), rs727504500, ClinGen CA183181, ClinVar RCV000155638, ClinVar RCV000766623, REVEL 0.39, CADD 25.70, Uncertain significance, not specified; not provided; Dilated cardiomyopathy 1C
- K68E (p.Lys68Glu), Ensembl rs1564633014
- K68N (p.Lys68Asn), TOPMed rs1844991986
- K68T (p.Lys68Thr), cosmic curated COSV10609, REVEL 0.54, CADD 27.90
- K68R (p.Lys68Arg), gnomAD 10-86679476-A-G, REVEL 0.32, CADD 27.40
- I69F (p.Ile69Phe), gnomAD rs1844992123, REVEL 0.58, CADD 29.00
- I69S (p.Ile69Ser), NCI-TCGA Cosmic COSV5393, cosmic curated COSV53937, TOPMed rs1844992241, Variant assessed as somatic; moderate impact.
- K70T (p.Lys70Thr), cosmic curated COSV53944
- K70Q (p.Lys70Gln), gnomAD 10-86679481-A-C, REVEL 0.47, CADD 27.00
- S71A (p.Ser71Ala), rs2492565035, ClinGen CA377451477, ClinVar RCV003054950, Uncertain significance, Myofibrillar myopathy 4
- S71C (p.Ser71Cys), rs772249948, ClinGen CA5584612, cosmic curated COSV53949, ClinVar RCV001765346, REVEL 0.25, CADD 26.10, Uncertain significance, Cardiovascular phenotype; not provided; Myofibrillar myopathy 4
- S71Y (p.Ser71Tyr), NCI-TCGA Cosmic COSV5394, Variant assessed as somatic; moderate impact.
- S71T (p.Ser71Thr), gnomAD 10-86679484-T-A, REVEL 0.09, CADD 25.30
- S71S (p.Ser71Ser), gnomAD 10-86679486-T-C, CADD 4.78
- A72V (p.Ala72Val), cosmic curated COSV99555, REVEL 0.32, CADD 26.70
- S73N (p.Ser73Asn), rs1844992525, ClinGen CA377451489, ClinVar RCV002613632, AlphaMissense 0.14, MetaLR 0.07, Uncertain significance, Myofibrillar myopathy 4
- S73T (p.Ser73Thr), rs1844992525, ClinGen CA377451490, ClinVar RCV001171120, Ensembl rs1844992525, REVEL 0.18, AlphaMissense 0.14, Uncertain significance, Cardiomyopathy
- N75I (p.Asn75Ile), gnomAD 10-86679497-A-T, REVEL 0.35, CADD 26.90
- N75S (p.Asn75Ser), gnomAD 10-86679497-A-G, REVEL 0.14, CADD 22.40
Public LDB3 analysis runs
- LDB3 analysis run — LDB3 (1,449 variants) — completed 2026-08-20