SFTPB (P07988) variants and mutations
SFTPB (also known as P07988) is a human protein-coding gene encoding a pulmonary surfactant-associated protein B protein. It lowers surface tension and stabilizes pulmonary surfactant films during repeated breathing cycles, preventing alveolar collapse at end expiration. Biallelic loss-of-function variants cause severe neonatal surfactant dysfunction and respiratory failure. This analysis covers 764 SFTPB variants and mutations. Of these, 76% have computational variant effect predictions. Disease context includes Neonatal acute respiratory distress with surfactant metabolism deficiency, surfactant metabolism dysfunction, pulmonary, 1, and Congenital pulmonary alveolar proteinosis. Example SFTPB variants include A2G, E3K, and S4L.
Variant analysis overview
- Gene: SFTPB
- Protein: P07988
- UniProt accession: P07988
- Organism: Homo sapiens
- Variants analyzed: 764
- Variant scope: all variants
- Completed: 2026-08-20
Variant and mutation evidence
- Variant composition: 544 unspecified-consequence records; 1 stop lost; 90 synonymous variants; 95 missense variants; 5 stop-gained variants; 15 frameshift variants; 5 splice-region variants; 4 in-frame deletions; 1 in-frame insertions; 3 substitution
- Prediction scores: 582 variants have prediction scores (76% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Neonatal acute respiratory distress with surfactant metabolism deficiency, surfactant metabolism dysfunction, pulmonary, 1, Congenital pulmonary alveolar proteinosis, hereditary pulmonary alveolar proteinosis, interstitial lung disease, newborn respiratory distress syndrome, respiratory distress syndrome in premature infants, Moderate albuminuria, alcohol drinking, acute respiratory distress syndrome, chronic obstructive pulmonary disease, non-small cell lung carcinoma.
Protein structure and variant hotspots
- Protein features: 4 domains; 2 post-translational modification sites.
- Structural context: 566 variants have structural context.
- PTM context: 4 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable SFTPB variants
Examples include A2G, E3K, S4L, H5P, H5Y, L7R, Q8R, W9*. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- A2G (p.Ala2Gly), TOPMed rs1297321720, gnomAD rs1297321720, REVEL 0.15, CADD 16.20
- E3K (p.Glu3Lys), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60894, REVEL 0.08, CADD 0.32, Variant assessed as somatic; moderate impact.
- S4L (p.Ser4Leu), gnomAD rs1359858876, REVEL 0.13, CADD 14.40
- H5P (p.His5Pro), Ensembl rs1573480844
- H5Y (p.His5Tyr), rs1427243362, ClinGen CA347493130, ClinVar RCV002223434, ClinVar RCV005742426, REVEL 0.07, CADD 6.86, Uncertain significance, Hereditary pulmonary alveolar proteinosis; not provided
- L7R (p.Leu7Arg), Ensembl rs1677752880
- Q8R (p.Gln8Arg), cosmic curated COSV60894, REVEL 0.12, CADD 0.02
- W9* (p.Trp9Ter), TOPMed rs1226457777, gnomAD rs1226457777, CADD 35.00
- W9L (p.Trp9Leu), TOPMed rs1226457777, gnomAD rs1226457777, REVEL 0.26, CADD 23.20
- W9R (p.Trp9Arg), gnomAD rs1164736987, REVEL 0.26, CADD 23.10
- L11P (p.Leu11Pro), rs886056385, ClinGen CA10616378, ClinVar RCV000379167, ClinVar RCV003168512, REVEL 0.57, CADD 23.10, Uncertain significance, Surfactant metabolism dysfunction, pulmonary, 1; Hereditary pulmonary alveolar p
- L11R (p.Leu11Arg), TOPMed rs886056385, gnomAD rs886056385, REVEL 0.59, CADD 24.40, Uncertain significance
- L11V (p.Leu11Val), Ensembl rs1573480797, REVEL 0.23, CADD 22.50
- L12R (p.Leu12Arg), gnomAD rs1184443469, REVEL 0.58, CADD 24.20
- L13P (p.Leu13Pro), TOPMed rs909160441, REVEL 0.69, CADD 24.30
- L14P (p.Leu14Pro), rs886056384, ClinGen CA10614546, ClinVar RCV000343248, ClinVar RCV006629136, REVEL 0.52, CADD 22.20, Uncertain significance, Surfactant metabolism dysfunction, pulmonary, 1; not provided
- P15T (p.Pro15Thr), gnomAD rs1250074206, REVEL 0.14, CADD 18.60
- T16M (p.Thr16Met), cosmic curated COSV10590, TOPMed rs1490852263, gnomAD rs1490852263, REVEL 0.08, CADD 2.02, Uncertain significance, not provided; Surfactant metabolism dysfunction, pulmonary, 1
- L17F (p.Leu17Phe), TOPMed rs1677748918, REVEL 0.11, CADD 15.70
- L17P (p.Leu17Pro), rs886056385, Uncertain significance
- C18Y (p.Cys18Tyr), TOPMed rs1294607351, gnomAD rs1294607351, REVEL 0.18, CADD 21.90
- G19C (p.Gly19Cys), TOPMed rs1358662762, gnomAD rs1358662762, REVEL 0.20, CADD 19.20
- G19D (p.Gly19Asp), TOPMed rs1367413630, gnomAD rs1367413630, REVEL 0.32, CADD 13.10
- G19R (p.Gly19Arg), TOPMed rs1358662762, gnomAD rs1358662762, REVEL 0.25, CADD 16.00
- P20Q (p.Pro20Gln), gnomAD rs1240915089, REVEL 0.24, CADD 12.50
- G21S (p.Gly21Ser), rs1677747290, ClinGen CA347493036, ClinVar RCV002387237, gnomAD rs1677747290, REVEL 0.06, CADD 10.30, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- A23D (p.Ala23Asp), gnomAD rs1403793073, REVEL 0.26, CADD 19.40
- A24S (p.Ala24Ser), TOPMed rs925336255, gnomAD rs925336255, REVEL 0.07, CADD 12.70
- A24T (p.Ala24Thr), rs925336255, TOPMed rs925336255, gnomAD rs925336255, REVEL 0.03, CADD 14.60, Variant assessed as somatic; moderate impact.
- W25* (p.Trp25Ter), ExAC rs763238120, TOPMed rs763238120, gnomAD rs763238120, cosmic curated COSV10742, CADD 34.00
- W25C (p.Trp25Cys), ExAC rs763238120, TOPMed rs763238120, gnomAD rs763238120, REVEL 0.15, CADD 17.40
- W25L (p.Trp25Leu), 1000Genomes rs561295206, ExAC rs561295206, gnomAD rs561295206, REVEL 0.10, CADD 12.80
- W25R (p.Trp25Arg), rs1320815322, NCI-TCGA Cosmic COSV6089, cosmic curated COSV60893, gnomAD rs1320815322, REVEL 0.09, CADD 0.00, Variant assessed as somatic; moderate impact.
- T27A (p.Thr27Ala), gnomAD rs1471042409, REVEL 0.07, CADD 0.06
- T27I (p.Thr27Ile), TOPMed rs1270553539, gnomAD rs1270553539, REVEL 0.07, CADD 14.80
- T27N (p.Thr27Asn), TOPMed rs1270553539, gnomAD rs1270553539, REVEL 0.09, CADD 13.60
- S29F (p.Ser29Phe), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60892, Variant assessed as somatic; moderate impact.
- S29Y (p.Ser29Tyr), TOPMed rs1443810880, gnomAD rs1443810880, REVEL 0.17, CADD 23.30, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- A31V (p.Ala31Val), ExAC rs765446107, TOPMed rs765446107, gnomAD rs765446107, REVEL 0.03, CADD 13.90
- A33D (p.Ala33Asp), cosmic curated COSV10819
- A33G (p.Ala33Gly), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60894, Variant assessed as somatic; moderate impact.
- A33T (p.Ala33Thr), Ensembl rs929248122
- Q34* (p.Gln34Ter), cosmic curated COSV10522
- Q34R (p.Gln34Arg), TOPMed rs922922988, gnomAD rs922922988, REVEL 0.03, CADD 9.01
- G35S (p.Gly35Ser), Ensembl rs1677729635, REVEL 0.78, CADD 25.20
- E37D (p.Glu37Asp), TOPMed rs1191122215, REVEL 0.07, CADD 18.40
- E37K (p.Glu37Lys), ExAC rs776744560, gnomAD rs776744560, REVEL 0.05, CADD 9.60
- F38L (p.Phe38Leu), cosmic curated COSV60893, gnomAD rs1195184532, NCI-TCGA Cosmic COSV6089, REVEL 0.39, CADD 27.00, Variant assessed as somatic; moderate impact.
- W39R (p.Trp39Arg), ExAC rs771970362, gnomAD rs771970362, REVEL 0.56, CADD 27.00
- Q41K (p.Gln41Lys), cosmic curated COSV10066
- S42I (p.Ser42Ile), cosmic curated COSV60894
- S42N (p.Ser42Asn), cosmic curated COSV60893
- L43P (p.Leu43Pro), TOPMed rs1247119186, gnomAD rs1247119186
- E44G (p.Glu44Gly), gnomAD rs1167954505, REVEL 0.36, CADD 27.90
- E44K (p.Glu44Lys), TOPMed rs979480452, gnomAD rs979480452, REVEL 0.28, CADD 25.80
- Q45* (p.Gln45Ter), rs1427648151, NCI-TCGA Cosmic COSV6089, cosmic curated COSV60894, TOPMed rs1427648151, AlphaMissense 0.09, MetaLR 0.14, Variant assessed as somatic; high impact.
- Q45E (p.Gln45Glu), TOPMed rs1427648151
- Q45K (p.Gln45Lys), rs1427648151, ClinGen CA347492784, ClinVar RCV004078508, AlphaMissense 0.09, MetaLR 0.14, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- A46E (p.Ala46Glu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A46S (p.Ala46Ser), rs774179232, ClinGen CA1744176, cosmic curated COSV60893, ClinVar RCV000377978, REVEL 0.59, CADD 23.90, Uncertain significance, Surfactant metabolism dysfunction, pulmonary, 1
- A46T (p.Ala46Thr), ExAC rs774179232, TOPMed rs774179232, gnomAD rs774179232, Uncertain significance
- Q48H (p.Gln48His), TOPMed rs1022876401, gnomAD rs1022876401
- Q48K (p.Gln48Lys), ExAC rs768442204, gnomAD rs768442204, REVEL 0.18, CADD 22.20
- C49Y (p.Cys49Tyr), rs1218322078, ClinGen CA347492727, ClinVar RCV002254437, gnomAD rs1218322078, REVEL 0.79, CADD 25.00, Pathogenic, not provided
- R50I (p.Arg50Ile), rs749043722, ClinGen CA1744174, ClinVar RCV002585380, ExAC rs749043722, REVEL 0.27, CADD 21.40, Uncertain significance, not provided
- R50K (p.Arg50Lys), cosmic curated COSV10819
- R50T (p.Arg50Thr), ExAC rs749043722, TOPMed rs749043722, gnomAD rs749043722, Uncertain significance
- A51G (p.Ala51Gly), Ensembl rs1573480186
- G53A (p.Gly53Ala), 1000Genomes rs543297835, TOPMed rs543297835, gnomAD rs543297835, REVEL 0.21, CADD 24.00, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- H54R (p.His54Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- C55Y (p.Cys55Tyr), ExAC rs779741450, gnomAD rs779741450, REVEL 0.80, CADD 24.90
- Q57H (p.Gln57His), cosmic curated COSV10819
- Q57P (p.Gln57Pro), gnomAD rs1677724066, REVEL 0.28, CADD 23.70
- E58D (p.Glu58Asp), cosmic curated COSV10819
- E58K (p.Glu58Lys), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60892, Variant assessed as somatic; moderate impact.
- E58Q (p.Glu58Gln), cosmic curated COSV10819
- V59A (p.Val59Ala), cosmic curated COSV10464, gnomAD rs1407364935, REVEL 0.36, CADD 23.50
- V59I (p.Val59Ile), gnomAD rs1454907306, REVEL 0.33, CADD 24.20
- H62R (p.His62Arg), gnomAD rs1677723407, REVEL 0.03, CADD 15.40
- V63A (p.Val63Ala), rs2466706948, ClinGen CA347492492, ClinVar RCV004455846, Likely benign, Hereditary pulmonary alveolar proteinosis
- V63L (p.Val63Leu), ExAC rs780804657, TOPMed rs780804657, gnomAD rs780804657, REVEL 0.08, CADD 14.80
- V63M (p.Val63Met), ExAC rs780804657, TOPMed rs780804657, gnomAD rs780804657, REVEL 0.14, CADD 17.50
- G64E (p.Gly64Glu), ExAC rs764512527, gnomAD rs764512527, REVEL 0.07, CADD 7.81
- G64R (p.Gly64Arg), rs148914290, ClinGen CA1744168, cosmic curated COSV60893, ClinVar RCV000894695, REVEL 0.11, CADD 15.80, Conflicting interpretations, not provided; Hereditary pulmonary alveolar proteinosis; Surfactant metabolism d
- A65=, NCI-TCGA TCGA novel, Variant assessed as somatic; low impact.
- L68V (p.Leu68Val), TOPMed rs1329909080, gnomAD rs1329909080, REVEL 0.49, CADD 23.00
- C69* (p.Cys69Ter), TOPMed rs1409485997, gnomAD rs1409485997, CADD 36.00
- E71* (p.Glu71Ter), cosmic curated COSV10066
- E71Q (p.Glu71Gln), gnomAD rs1348659421, REVEL 0.43, CADD 23.70
- E71V (p.Glu71Val), gnomAD rs1305048454
- C72* (p.Cys72Ter), cosmic curated COSV10742, CADD 23.10
- E73K (p.Glu73Lys), 1000Genomes rs541110574, ExAC rs541110574, TOPMed rs541110574, gnomAD rs541110574, REVEL 0.30, CADD 13.30
- D74N (p.Asp74Asn), TOPMed rs1018017556, gnomAD rs1018017556, REVEL 0.22, CADD 16.50, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- V76I (p.Val76Ile), rs753519344, ClinGen CA1744132, NCI-TCGA Cosmic COSV1006, cosmic curated COSV10066, REVEL 0.14, CADD 5.47, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- H77R (p.His77Arg), TOPMed rs1479926793
- L79F (p.Leu79Phe), TOPMed rs761090575
- L79I (p.Leu79Ile), TOPMed rs761090575
- K81T (p.Lys81Thr), NCI-TCGA Cosmic COSV1006, cosmic curated COSV10066, Variant assessed as somatic; moderate impact.
- M82I (p.Met82Ile), gnomAD rs1677689390, REVEL 0.38, CADD 21.20
- A83S (p.Ala83Ser), 1000Genomes rs573709240, ExAC rs573709240, gnomAD rs573709240, REVEL 0.45, CADD 18.70
- A83T (p.Ala83Thr), 1000Genomes rs573709240, ExAC rs573709240, gnomAD rs573709240, REVEL 0.23, CADD 13.20, Likely benign, Hereditary pulmonary alveolar proteinosis
- E85K (p.Glu85Lys), cosmic curated COSV10464, REVEL 0.45, CADD 24.70
- E85V (p.Glu85Val), Ensembl rs2104416841
- A86V (p.Ala86Val), gnomAD rs1248908375, REVEL 0.27, CADD 14.10
- I87T (p.Ile87Thr), TOPMed rs1677688226
- I87V (p.Ile87Val), gnomAD rs1200961574, REVEL 0.24, CADD 15.10
- F88L (p.Phe88Leu), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60894, Ensembl rs981012857, REVEL 0.47, CADD 23.20, Variant assessed as somatic; moderate impact.
- Q89R (p.Gln89Arg), gnomAD rs1677687817, REVEL 0.62, CADD 32.00
- D90N (p.Asp90Asn), rs1248137913, NCI-TCGA Cosmic COSV1006, cosmic curated COSV10066, TOPMed rs1248137913, REVEL 0.23, CADD 16.50, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- T91K (p.Thr91Lys), rs45488101, ClinGen CA1744105, ClinVar RCV003559025, 1000Genomes rs45488101, REVEL 0.37, CADD 0.23, Uncertain significance, not provided
- T91M (p.Thr91Met), rs45488101, ClinGen CA1744104, cosmic curated COSV60893, ClinVar RCV002325780, REVEL 0.39, CADD 0.32, Conflicting interpretations, Hereditary pulmonary alveolar proteinosis; not provided
- M92I (p.Met92Ile), cosmic curated COSV60893
- M92T (p.Met92Thr), ExAC rs757279120, gnomAD rs757279120, REVEL 0.50, CADD 5.97
- R93K (p.Arg93Lys), TOPMed rs1677667354, REVEL 0.17, CADD 1.12
- K94N (p.Lys94Asn), ExAC rs751745613, TOPMed rs751745613, gnomAD rs751745613, REVEL 0.14, CADD 13.60, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- L96P (p.Leu96Pro), ExAC rs765241667
- E97D (p.Glu97Asp), 1000Genomes rs34682912, ESP rs34682912, ExAC rs34682912, TOPMed rs34682912, Benign
- E97G (p.Glu97Gly), ExAC rs755008142, TOPMed rs755008142, gnomAD rs755008142, REVEL 0.39, CADD 22.40, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- Q98* (p.Gln98Ter), 1000Genomes rs564056875, TOPMed rs564056875
- Q98E (p.Gln98Glu), 1000Genomes rs564056875, TOPMed rs564056875, REVEL 0.14, CADD 8.13
- Q98H (p.Gln98His), ExAC rs766040982, TOPMed rs766040982, gnomAD rs766040982
- Q98K (p.Gln98Lys), cosmic curated COSV60893
- E99D (p.Glu99Asp), 1000Genomes rs189048961, ExAC rs189048961, TOPMed rs189048961, gnomAD rs189048961, REVEL 0.16, CADD 8.27
- E99K (p.Glu99Lys), TOPMed rs1351865587, gnomAD rs1351865587, REVEL 0.49, CADD 17.30
- N101K (p.Asn101Lys), ExAC rs772677222, TOPMed rs772677222, gnomAD rs772677222, REVEL 0.11, CADD 0.03, Likely benign
- V102I (p.Val102Ile), rs767270671, ClinGen CA1744095, cosmic curated COSV60894, ClinVar RCV004305672, REVEL 0.23, CADD 0.00, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- V102L (p.Val102Leu), rs767270671, ClinGen CA347491303, ClinVar RCV001139493, ClinVar RCV004659360, REVEL 0.19, CADD 0.00, Uncertain significance, Surfactant metabolism dysfunction, pulmonary, 1; Hereditary pulmonary alveolar p
- P104S (p.Pro104Ser), gnomAD rs1245393843, REVEL 0.65, CADD 23.70
- K106E (p.Lys106Glu), TOPMed rs1349297564, REVEL 0.43, CADD 25.10
- K106R (p.Lys106Arg), TOPMed rs1677663668, REVEL 0.47, CADD 23.40, Uncertain significance, not provided
- L108F (p.Leu108Phe), cosmic curated COSV60893, REVEL 0.27, CADD 17.70
- L108P (p.Leu108Pro), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- M109V (p.Met109Val), cosmic curated COSV60892, ExAC rs773902434, gnomAD rs773902434, REVEL 0.22, CADD 3.85
- P110L (p.Pro110Leu), NCI-TCGA TCGA novel, TOPMed rs1677662851, Variant assessed as somatic; moderate impact.
- P110S (p.Pro110Ser), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60892, REVEL 0.10, CADD 16.20, Variant assessed as somatic; moderate impact.
- Q111H (p.Gln111His), TOPMed rs1280741950, gnomAD rs1280741950, REVEL 0.21, CADD 16.00
- C112* (p.Cys112Ter), gnomAD rs1298213949, CADD 33.00
- C112G (p.Cys112Gly), TOPMed rs1224230169, gnomAD rs1224230169, REVEL 0.79, CADD 24.20
- C112Y (p.Cys112Tyr), ExAC rs768183539, gnomAD rs768183539, REVEL 0.81, CADD 23.70
- Q114* (p.Gln114Ter), TOPMed rs1677661711
- V115M (p.Val115Met), gnomAD rs1329039539, REVEL 0.16, CADD 0.09
- D117E (p.Asp117Glu), ESP rs147417469, ExAC rs147417469, TOPMed rs147417469, gnomAD rs147417469, REVEL 0.15, CADD 2.13, Likely benign
- D117H (p.Asp117His), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60894, Variant assessed as somatic; moderate impact.
- D118E (p.Asp118Glu), Ensembl rs2104415166, REVEL 0.06, CADD 5.57
- D118G (p.Asp118Gly), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- D118N (p.Asp118Asn), rs45557339, ClinGen CA1744090, cosmic curated COSV60892, ClinVar RCV000758242, REVEL 0.06, CADD 0.03, Uncertain significance, not provided; Surfactant metabolism dysfunction, pulmonary, 1; Hereditary pulmon
- D118Y (p.Asp118Tyr), 1000Genomes rs45557339, ESP rs45557339, ExAC rs45557339, TOPMed rs45557339, REVEL 0.38, CADD 2.10, Uncertain significance
- Y119* (p.Tyr119Ter), ESP rs368293273, ExAC rs368293273, TOPMed rs368293273, gnomAD rs368293273, Likely benign
- Y119C (p.Tyr119Cys), cosmic curated COSV10888, Ensembl rs1677660901
- Y119N (p.Tyr119Asn), Ensembl rs2104415151
- F120L (p.Phe120Leu), rs138729391, ClinGen CA1744088, ClinVar RCV003815103, ESP rs138729391, REVEL 0.11, CADD 8.64, Uncertain significance, not provided
- F120S (p.Phe120Ser), TOPMed rs1401046724, gnomAD rs1401046724, REVEL 0.41, CADD 23.00
- F120V (p.Phe120Val), ESP rs138729391, ExAC rs138729391, TOPMed rs138729391, gnomAD rs138729391, Uncertain significance
- P121A (p.Pro121Ala), rs141905538, ClinGen CA1744087, ClinVar RCV001139492, ClinVar RCV003163307, REVEL 0.39, CADD 20.40, Conflicting interpretations, Surfactant metabolism dysfunction, pulmonary, 1; Hereditary pulmonary alveolar p
- P121S (p.Pro121Ser), ExAC rs141905538, TOPMed rs141905538, gnomAD rs141905538, REVEL 0.31, CADD 16.70, Uncertain significance
- P121T (p.Pro121Thr), ExAC rs141905538, TOPMed rs141905538, gnomAD rs141905538, REVEL 0.44, CADD 20.90, Uncertain significance
- P121X, rs779795223, Pathogenic
- L122P (p.Leu122Pro), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- L122R (p.Leu122Arg), rs1677658252, ClinGen CA1266878774, ClinVar RCV000014089, ClinVar RCV002513036, Pathogenic
- V123A (p.Val123Ala), TOPMed rs1677658104, REVEL 0.37, CADD 21.00
- I124V (p.Ile124Val), rs2466699768, ClinGen CA347491002, ClinVar RCV002321448, REVEL 0.17, CADD 1.52, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- D125N (p.Asp125Asn), rs140667432, ClinGen CA1744084, ClinVar RCV001139491, 1000Genomes rs140667432, REVEL 0.14, CADD 11.70, Uncertain significance, Surfactant metabolism dysfunction, pulmonary, 1
- Y126D (p.Tyr126Asp), rs184305471, ClinGen CA1744082, cosmic curated COSV60892, ClinVar RCV001139490, REVEL 0.51, CADD 24.80, Uncertain significance, Surfactant metabolism dysfunction, pulmonary, 1; Hereditary pulmonary alveolar p
- Y126H (p.Tyr126His), 1000Genomes rs184305471, ExAC rs184305471, TOPMed rs184305471, gnomAD rs184305471, REVEL 0.10, CADD 21.20, Uncertain significance
- F127C (p.Phe127Cys), gnomAD rs1677657202, REVEL 0.59, CADD 26.60
- N129I (p.Asn129Ile), Ensembl rs1416151726, REVEL 0.18, CADD 19.80
- N129K (p.Asn129Lys), ExAC rs758573590, TOPMed rs758573590, gnomAD rs758573590, cosmic curated COSV60893, REVEL 0.13, CADD 14.60
- Q130E (p.Gln130Glu), ExAC rs753771008, gnomAD rs753771008, REVEL 0.22, CADD 18.80
- Q130H (p.Gln130His), Ensembl rs879101334
- Q130L (p.Gln130Leu), gnomAD rs1677656392, REVEL 0.34, CADD 23.00
- Q130R (p.Gln130Arg), NCI-TCGA Cosmic COSV6089, cosmic curated COSV60893, REVEL 0.27, CADD 23.90, Variant assessed as somatic; moderate impact.
- T131I (p.Thr131Ile), rs1130866, ClinGen CA177942, cosmic curated COSV60892, ClinVar RCV000151850, REVEL 0.15, CADD 15.50, Benign, Hereditary pulmonary alveolar proteinosis; not specified; not provided
- T131S (p.Thr131Ser), 1000Genomes rs1130866, ESP rs1130866, ExAC rs1130866, TOPMed rs1130866, REVEL 0.21, CADD 22.80, Benign
- D132=, rs529554098, NCI-TCGA Cosmic COSV6089, Variant assessed as somatic; low impact.
- D132N (p.Asp132Asn), gnomAD rs1378315214
- G135S (p.Gly135Ser), rs35373464, ClinGen CA1744041, cosmic curated COSV10522, ClinVar RCV000728151, REVEL 0.36, CADD 9.13, Conflicting interpretations, not provided; Surfactant metabolism dysfunction, pulmonary, 1; Hereditary pulmon
- G135V (p.Gly135Val), rs1289542876, NCI-TCGA Cosmic COSV1006, cosmic curated COSV10066, gnomAD rs1289542876, REVEL 0.17, CADD 0.75, Variant assessed as somatic; moderate impact.
- I136N (p.Ile136Asn), rs1210349465, ClinGen CA347490758, ClinVar RCV002328269, TOPMed rs1210349465, REVEL 0.61, CADD 24.40, Uncertain significance, Hereditary pulmonary alveolar proteinosis
- M138T (p.Met138Thr), rs777381019, ClinGen CA1744039, ClinVar RCV001137242, ExAC rs777381019, REVEL 0.09, CADD 1.63, Uncertain significance, Surfactant metabolism dysfunction, pulmonary, 1
- M138V (p.Met138Val), ExAC rs751412409, gnomAD rs751412409, REVEL 0.12, CADD 0.28
Public SFTPB analysis runs
- SFTPB analysis run — SFTPB (764 variants) — completed 2026-08-20