RP2 (Protein XRP2) variants and mutations
RP2 (also known as Protein XRP2) is a human protein-coding gene encoding a protein XRP2 protein. It regulates small-GTPase and ciliary trafficking processes required for photoreceptor maintenance. Loss-of-function variants cause X-linked retinitis pigmentosa, often with early-onset and severe rod-cone degeneration. This analysis covers 661 RP2 variants and mutations. Of these, 82% have computational variant effect predictions. Disease context includes retinitis pigmentosa, retinitis pigmentosa 2, and Retinal dystrophy. Example RP2 variants include M1K, M1L, and M1R.
Variant analysis overview
- Gene: RP2
- Protein: Protein XRP2
- UniProt accession: O75695
- Organism: Homo sapiens
- Variants analyzed: 661
- Variant scope: all variants
- Completed: 2026-08-22
Variant and mutation evidence
- Variant composition: 348 unspecified-consequence records; 180 missense variants; 8 stop-gained variants; 103 synonymous variants; 14 frameshift variants; 3 in-frame deletions; 4 splice-region variants; 3 stop lost; 1 substitution
- Prediction scores: 544 variants have prediction scores (82% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: retinitis pigmentosa, retinitis pigmentosa 2, Retinal dystrophy, retinitis pigmentosa 3, Leber congenital amaurosis, retinal disorder, eye disorder, RP2-related retinopathy, Cone rod dystrophy, cone-rod dystrophy, Macular dystrophy, Abnormality of the eye.
Protein structure and variant hotspots
- Protein features: 1 domains; 2 binding sites.
- Structural context: 258 variants have structural context.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable RP2 variants
Examples include M1K, M1L, M1R, M1T, M1V, G2C, G2S, G2D. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1K (p.Met1Lys), rs797044561, ClinGen CA413038134, ClinVar RCV001902474, MetaLR 0.84, MetaSVM 0.76, Pathogenic, not provided
- M1L (p.Met1Leu), rs2147074594, ClinGen CA413038133, ClinVar RCV003006391, ClinVar RCV005254661, MetaLR 0.84, MetaSVM 0.76, Pathogenic/Likely pathogenic, Retinitis pigmentosa 2; not provided
- M1R (p.Met1Arg), rs797044561, ClinGen CA413038135, ClinVar RCV002824425, MetaLR 0.84, MetaSVM 0.76, Pathogenic, not provided
- M1T (p.Met1Thr), rs797044561, ClinGen CA236346, ClinVar RCV000171435, ClinVar RCV001003180, MetaLR 0.84, MetaSVM 0.76, Pathogenic
- M1V (p.Met1Val), rs2147074594, ClinGen CA413038132, ClinVar RCV001946602, MetaLR 0.84, MetaSVM 0.76, Pathogenic, not provided
- G2C (p.Gly2Cys), rs1556313408, ClinGen CA413038141, ClinVar RCV003044991, AlphaMissense 0.64, MetaLR 0.87, Uncertain significance, not provided
- G2S (p.Gly2Ser), rs1556313408, ClinGen CA413038139, ClinVar RCV002819618, gnomAD rs1556313408, REVEL 0.72, AlphaMissense 0.64, Uncertain significance, not provided
- G2D (p.Gly2Asp), gnomAD X-46837105-G-A, REVEL 0.77, CADD 26.40
- G2V (p.Gly2Val), gnomAD X-46837105-G-T, REVEL 0.89, CADD 26.30
- C3G (p.Cys3Gly), Ensembl rs917893829
- C3S (p.Cys3Ser), rs782344765, ClinGen CA10394159, ClinVar RCV000479201, ClinVar RCV002470866, REVEL 0.86, CADD 26.20, Conflicting interpretations, Retinal dystrophy; not provided; Retinitis pigmentosa 2
- C3F (p.Cys3Phe), gnomAD X-46837108-G-T, REVEL 0.80, CADD 27.30
- C3Y (p.Cys3Tyr), gnomAD X-46837108-G-A, REVEL 0.80, CADD 27.10
- C3* (p.Cys3Ter), gnomAD X-46837109-C-A, CADD 34.00
- F4* (p.Phe4Ter), rs2147074613, ClinGen CA2573158910, ClinVar RCV001946613, Ensembl rs2147074613, Pathogenic
- F4C (p.Phe4Cys), rs782190396, ClinGen CA10394160, ClinVar RCV001168266, ClinVar RCV001522598, REVEL 0.23, CADD 21.80, Conflicting interpretations, not provided; Retinitis pigmentosa
- F4L (p.Phe4Leu), gnomAD X-46837112-C-A, REVEL 0.24, CADD 20.30
- F5S (p.Phe5Ser), gnomAD X-46837114-T-C, REVEL 0.56, CADD 23.50
- S6C (p.Ser6Cys), gnomAD rs1556313431, REVEL 0.41, CADD 23.20
- S6F (p.Ser6Phe), gnomAD X-46837117-C-T, REVEL 0.43, CADD 23.50
- S6Y (p.Ser6Tyr), gnomAD X-46837117-C-A, REVEL 0.57, CADD 24.70
- S6S (p.Ser6Ser), gnomAD X-46837118-C-A, CADD 13.50
- K7Q (p.Lys7Gln), rs1924520196, ClinGen CA413038172, ClinVar RCV001074934, ClinVar RCV001862583, REVEL 0.45, CADD 26.40, Uncertain significance, not provided; Retinal dystrophy
- K7R (p.Lys7Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- K7E (p.Lys7Glu), gnomAD X-46837119-A-G, REVEL 0.47, CADD 26.60
- K7N (p.Lys7Asn), gnomAD X-46837121-G-T, REVEL 0.38, CADD 25.50
- R8* (p.Arg8Ter), rs2147074627, ClinGen CA413038181, ClinVar RCV001956114, Ensembl rs2147074627, CADD 35.00, Pathogenic
- R8K (p.Arg8Lys), gnomAD X-46837123-G-A, REVEL 0.21, CADD 15.20
- R8I (p.Arg8Ile), gnomAD X-46837123-G-T, REVEL 0.26, CADD 17.60
- R9L (p.Arg9Leu), TOPMed rs1351349465, gnomAD rs1351349465, REVEL 0.26, CADD 19.60
- R9W (p.Arg9Trp), TOPMed rs1206639289, gnomAD rs1206639289, REVEL 0.34, CADD 23.50
- R9Q (p.Arg9Gln), gnomAD X-46837126-G-A, REVEL 0.20, CADD 19.40
- R9R (p.Arg9Arg), rs1556313439, gnomAD X-46837127-G-A, CADD 14.60
- K10* (p.Lys10Ter), rs1556313447, ClinGen CA413038194, ClinVar RCV003890471, AlphaMissense 0.09, MetaLR 0.49, Likely pathogenic
- K10E (p.Lys10Glu), rs1556313447, ClinGen CA413038193, ClinVar RCV002223739, gnomAD rs1556313447, REVEL 0.41, AlphaMissense 0.09, Uncertain significance, not provided
- K10N (p.Lys10Asn), gnomAD X-46837130-G-T, REVEL 0.30, CADD 19.70
- K10K (p.Lys10Lys), rs782402689, gnomAD X-46837130-G-A, CADD 13.40
- A11V (p.Ala11Val), gnomAD X-46837132-C-T, REVEL 0.15, CADD 15.50
- A11D (p.Ala11Asp), gnomAD X-46837132-C-A, REVEL 0.11, CADD 13.80
- D12G (p.Asp12Gly), gnomAD rs1556313463, REVEL 0.18, CADD 12.60
- D12N (p.Asp12Asn), gnomAD X-46837134-G-A, REVEL 0.19, CADD 17.80
- D12Y (p.Asp12Tyr), gnomAD X-46837134-G-T, REVEL 0.21, CADD 22.40
- D12V (p.Asp12Val), gnomAD X-46837135-A-T, REVEL 0.20, CADD 12.80
- K13* (p.Lys13Ter), rs1924521211, ClinGen CA413038216, ClinVar RCV001074570, Ensembl rs1924521211, Likely pathogenic
- K13M (p.Lys13Met), rs1238437293, ClinGen CA413038219, ClinVar RCV001075679, TOPMed rs1238437293, REVEL 0.24, CADD 17.60, Uncertain significance, Retinal dystrophy
- K13E (p.Lys13Glu), gnomAD X-46837137-A-G, REVEL 0.26, CADD 16.60
- K13R (p.Lys13Arg), gnomAD X-46837138-A-G, REVEL 0.13, CADD 15.10
- K13K (p.Lys13Lys), gnomAD X-46837139-G-A, CADD 10.30
- E14* (p.Glu14Ter), gnomAD X-46837140-G-T, CADD 35.00
- E14D (p.Glu14Asp), gnomAD X-46837142-G-T, REVEL 0.21, CADD 10.70
- E14E (p.Glu14Glu), gnomAD X-46837142-G-A, CADD 8.36
- S15L (p.Ser15Leu), rs1556313479, ClinGen CA413038235, NCI-TCGA Cosmic COSV5446, ClinVar RCV001321622, REVEL 0.14, CADD 19.00, Uncertain significance, Retinal dystrophy; not provided
- S15W (p.Ser15Trp), NCI-TCGA Cosmic COSV5446, TOPMed rs1556313479, gnomAD rs1556313479, REVEL 0.33, CADD 22.80, Uncertain significance, Stargardt disease
- S15R (p.Ser15Arg), rs1556313474, gnomAD X-46837142-GT-G, CADD 22.30
- S15* (p.Ser15Ter), gnomAD X-46837144-C-A, CADD 34.00
- S15S (p.Ser15Ser), gnomAD X-46837145-G-A, CADD 11.40
- R16L (p.Arg16Leu), rs782026786, ClinGen CA413038238, ClinVar RCV003355160, ClinVar RCV003549077, REVEL 0.15, CADD 12.90, Uncertain significance, not provided; Inborn genetic diseases
- R16P (p.Arg16Pro), ExAC rs782026786, TOPMed rs782026786, gnomAD rs782026786, REVEL 0.10, CADD 13.50
- R16Q (p.Arg16Gln), ExAC rs782026786, TOPMed rs782026786, gnomAD rs782026786, REVEL 0.18, CADD 12.50
- R16W (p.Arg16Trp), NCI-TCGA Cosmic COSV5446, REVEL 0.15, CADD 19.50, Variant assessed as somatic; moderate impact.
- R16R (p.Arg16Arg), gnomAD X-46837146-C-A, CADD 9.14
- P17L (p.Pro17Leu), rs782387061, ClinGen CA10394164, ClinVar RCV000416240, ClinVar RCV003362778, REVEL 0.20, CADD 13.90, Conflicting interpretations, Inborn genetic diseases; not provided
- P17R (p.Pro17Arg), rs782387061, ClinGen CA10394165, ClinVar RCV002650076, ExAC rs782387061, REVEL 0.20, CADD 12.60, Uncertain significance, not provided
- P17S (p.Pro17Ser), rs782103396, ClinGen CA10394163, ClinVar RCV000787703, ClinVar RCV001797794, REVEL 0.24, CADD 1.21, Conflicting interpretations, not specified; not provided; Retinitis pigmentosa 2
- P17T (p.Pro17Thr), gnomAD X-46837149-C-A, REVEL 0.22, CADD 0.78
- P17H (p.Pro17His), gnomAD X-46837150-C-A, REVEL 0.27, CADD 14.50
- P17P (p.Pro17Pro), rs370530958, gnomAD X-46837151-C-T, CADD 7.74
- E18K (p.Glu18Lys), ExAC rs782717555, TOPMed rs782717555, gnomAD rs782717555, REVEL 0.12, CADD 12.70
- E18* (p.Glu18Ter), gnomAD X-46837152-G-T, CADD 31.00
- E18V (p.Glu18Val), gnomAD X-46837153-A-T, REVEL 0.19, CADD 16.60
- E18G (p.Glu18Gly), gnomAD X-46837153-A-G, REVEL 0.17, CADD 16.70
- E18D (p.Glu18Asp), gnomAD X-46837154-G-T, REVEL 0.20, CADD 11.70
- E18E (p.Glu18Glu), gnomAD X-46837154-G-A, CADD 8.47
- N19K (p.Asn19Lys), rs1924523153, ClinGen CA413038256, ClinVar RCV001341652, Ensembl rs1924523153, REVEL 0.25, CADD 7.32, Uncertain significance, not provided
- N19S (p.Asn19Ser), TOPMed rs1924523013, REVEL 0.25, CADD 3.68
- N19R (p.Asn19Arg), gnomAD X-46837150-CCG-C, CADD 20.40
- N19N (p.Asn19Asn), gnomAD X-46837157-C-T, CADD 8.50
- E20* (p.Glu20Ter), rs1924523272, ClinGen CA413038259, ClinVar RCV001382693, ClinVar RCV005438985, CADD 29.10, Pathogenic
- E20G (p.Glu20Gly), Ensembl rs1924523547, REVEL 0.14, CADD 18.40
- E20K (p.Glu20Lys), Ensembl rs1924523272, REVEL 0.21, CADD 9.48, Pathogenic
- E20E (p.Glu20Glu), gnomAD X-46837160-G-A, CADD 8.86
- E20D (p.Glu20Asp), gnomAD X-46837160-G-T, REVEL 0.17, CADD 11.40
- E21* (p.Glu21Ter), gnomAD X-46837161-G-T, CADD 34.00
- E21K (p.Glu21Lys), gnomAD X-46837161-G-A, REVEL 0.20, CADD 20.50
- E21E (p.Glu21Glu), gnomAD X-46837163-G-A, CADD 10.10
- E21D (p.Glu21Asp), gnomAD X-46837163-G-T, REVEL 0.14, CADD 16.30
- E22D (p.Glu22Asp), TOPMed rs1924523700, REVEL 0.22, CADD 15.10, Uncertain significance, not provided
- E22del (p.Glu22del), rs1556313506, gnomAD X-46837157-CGAG-C, CADD 14.60
- E22K (p.Glu22Lys), gnomAD X-46837164-G-A, REVEL 0.27, CADD 20.70
- E22* (p.Glu22Ter), gnomAD X-46837164-G-T, CADD 34.00
- E22G (p.Glu22Gly), gnomAD X-46837165-A-G, REVEL 0.21, CADD 22.60
- E22E (p.Glu22Glu), gnomAD X-46837166-G-A, CADD 9.54
- R23Q (p.Arg23Gln), rs782167265, ClinGen CA10394169, ClinVar RCV002020025, ExAC rs782167265, REVEL 0.18, CADD 0.13, Uncertain significance, not provided
- R23W (p.Arg23Trp), rs200053312, ClinGen CA10394168, ClinVar RCV001983209, ClinVar RCV003250351, REVEL 0.18, CADD 22.50, Uncertain significance, Inborn genetic diseases; not provided
- R23R (p.Arg23Arg), gnomAD X-46837167-C-A, CADD 11.20
- R23P (p.Arg23Pro), gnomAD X-46837168-G-C, REVEL 0.15, CADD 0.36
- R23L (p.Arg23Leu), gnomAD X-46837168-G-T, REVEL 0.21, CADD 0.25
- P24L (p.Pro24Leu), rs2147074680, ClinGen CA413038295, ClinVar RCV001974036, Ensembl rs2147074680, REVEL 0.37, CADD 20.60, Uncertain significance, not provided
- P24S (p.Pro24Ser), gnomAD X-46837170-C-T, REVEL 0.28, CADD 22.40
- P24T (p.Pro24Thr), gnomAD X-46837170-C-A, REVEL 0.34, CADD 18.40
- P24Q (p.Pro24Gln), gnomAD X-46837171-C-A, REVEL 0.32, CADD 18.70
- P24P (p.Pro24Pro), rs1556313519, gnomAD X-46837172-A-C, CADD 7.84
- K25T (p.Lys25Thr), rs1556313523, ClinGen CA413038299, ClinVar RCV003679696, gnomAD rs1556313523, REVEL 0.48, CADD 25.20, Uncertain significance, not provided
- K25R (p.Lys25Arg), gnomAD X-46837174-A-G, REVEL 0.31, CADD 22.40
- K25M (p.Lys25Met), gnomAD X-46837174-A-T, REVEL 0.48, CADD 23.90
- K25N (p.Lys25Asn), gnomAD X-46837175-G-T, REVEL 0.37, CADD 22.80
- K25K (p.Lys25Lys), gnomAD X-46837175-G-A, CADD 12.70
- Q26* (p.Gln26Ter), rs104894925, ClinGen CA255299, ClinVar RCV000011291, ClinVar RCV000657655, CADD 35.00, Pathogenic
- Q26K (p.Gln26Lys), gnomAD X-46837176-C-A, REVEL 0.27, CADD 15.90
- Q26Q (p.Gln26Gln), gnomAD X-46837178-G-A, CADD 13.40
- Q26H (p.Gln26His), gnomAD X-46837178-G-T, REVEL 0.39, CADD 23.30
- Y27* (p.Tyr27Ter), rs2519902152, ClinGen CA2580100999, ClinVar RCV003022633, CADD 35.00, Pathogenic
- Y27N (p.Tyr27Asn), gnomAD X-46837179-T-A, REVEL 0.63, CADD 27.60
- S28G (p.Ser28Gly), gnomAD X-46837182-A-G, REVEL 0.52, CADD 26.70
- S28C (p.Ser28Cys), gnomAD X-46837182-A-T, REVEL 0.67, CADD 27.40
- S28N (p.Ser28Asn), gnomAD X-46837183-G-A, REVEL 0.48, CADD 26.90
- S28I (p.Ser28Ile), gnomAD X-46837183-G-T, REVEL 0.68, CADD 28.60
- S28S (p.Ser28Ser), gnomAD X-46837184-C-T, CADD 15.70
- S28R (p.Ser28Arg), gnomAD X-46837184-C-A, REVEL 0.62, CADD 27.30
- W29* (p.Trp29Ter), rs2147074689, ClinGen CA413038343, ClinVar RCV001946850, ClinVar RCV003888942, CADD 37.00, Pathogenic
- W29R (p.Trp29Arg), gnomAD X-46837185-T-C, REVEL 0.60, CADD 31.00
- W29L (p.Trp29Leu), gnomAD X-46837186-G-T, REVEL 0.56, CADD 28.60
- W29C (p.Trp29Cys), gnomAD X-46837187-G-T, REVEL 0.63, CADD 31.00
- D30G (p.Asp30Gly), TOPMed rs1386345335, gnomAD rs1386345335, REVEL 0.60, CADD 25.50, Uncertain significance, not provided
- D30H (p.Asp30His), ESP rs377324837, ExAC rs377324837, gnomAD rs377324837, REVEL 0.57, CADD 28.50
- D30Y (p.Asp30Tyr), NCI-TCGA Cosmic COSV5446, REVEL 0.73, CADD 29.10, Variant assessed as somatic; moderate impact.
- Q31* (p.Gln31Ter), rs2147074694, ClinGen CA413038359, ClinVar RCV001389355, Ensembl rs2147074694, Pathogenic
- Q31H (p.Gln31His), gnomAD rs1556313543, REVEL 0.22, CADD 22.60
- Q31R (p.Gln31Arg), gnomAD X-46837192-A-G, REVEL 0.31, CADD 22.60
- Q31Q (p.Gln31Gln), rs1556313543, gnomAD X-46837193-G-A, CADD 12.80
- R32L (p.Arg32Leu), rs781872752, ClinGen CA10394171, ClinVar RCV003842172, ExAC rs781872752, REVEL 0.68, CADD 29.30, Benign, not provided
- R32S (p.Arg32Ser), gnomAD X-46837194-C-A, REVEL 0.66, CADD 26.60
- R32C (p.Arg32Cys), gnomAD X-46837194-C-T, REVEL 0.70, CADD 32.00
- R32R (p.Arg32Arg), gnomAD X-46837196-C-A, CADD 12.40
- E33K (p.Glu33Lys), NCI-TCGA TCGA novel, REVEL 0.21, CADD 22.00, Variant assessed as somatic; moderate impact.
- E33* (p.Glu33Ter), gnomAD X-46837197-G-T, CADD 35.00
- E33D (p.Glu33Asp), gnomAD X-46837199-G-T, REVEL 0.22, CADD 17.70
- K34E (p.Lys34Glu), rs782473693, ClinGen CA10394172, ClinVar RCV001347539, ClinVar RCV004758791, REVEL 0.50, CADD 23.40, Uncertain significance, not provided
- K34R (p.Lys34Arg), gnomAD X-46837201-A-G, REVEL 0.31, CADD 25.10
- V35I (p.Val35Ile), ExAC rs782634392, gnomAD rs782634392, REVEL 0.32, CADD 15.80
- V35L (p.Val35Leu), gnomAD X-46853476-G-C, REVEL 0.26, CADD 20.20
- P37A (p.Pro37Ala), gnomAD X-46853482-C-G, REVEL 0.32, CADD 15.00
- D39N (p.Asp39Asn), gnomAD X-46853488-G-A, REVEL 0.52, CADD 22.80
- D39V (p.Asp39Val), gnomAD X-46853489-A-T, REVEL 0.83, CADD 25.70
- Y40C (p.Tyr40Cys), TOPMed rs1924894872, gnomAD rs1924894872, REVEL 0.79, CADD 24.60, Uncertain significance, Inborn genetic diseases
- Y40D (p.Tyr40Asp), gnomAD X-46853491-T-G, REVEL 0.87, CADD 26.40
- M41I (p.Met41Ile), rs145720330, ClinGen CA10394182, ClinVar RCV001511504, ESP rs145720330, REVEL 0.25, CADD 14.30, Benign, not provided
- M41T (p.Met41Thr), rs782356034, ClinGen CA10394181, ClinVar RCV001237870, ExAC rs782356034, REVEL 0.29, CADD 12.00, Likely benign, not provided
- M41V (p.Met41Val), rs141869514, ClinGen CA10394180, ClinVar RCV001917570, ESP rs141869514, REVEL 0.28, CADD 16.50, Benign, not provided
- F42L (p.Phe42Leu), NCI-TCGA Cosmic COSV5446, ExAC rs782287231, TOPMed rs782287231, REVEL 0.21, CADD 17.60, Uncertain significance, not provided
- S43G (p.Ser43Gly), rs201111874, ClinGen CA10394184, ClinVar RCV001201464, ClinVar RCV003890343, REVEL 0.34, CADD 19.20, Uncertain significance, not provided; Retinal dystrophy
- G44* (p.Gly44Ter), NCI-TCGA Cosmic COSV5446, Variant assessed as somatic; high impact.
- G44E (p.Gly44Glu), TOPMed rs1556318533, gnomAD rs1556318533, REVEL 0.49, CADD 21.30
- K46R (p.Lys46Arg), Ensembl rs1924895872
- D47G (p.Asp47Gly), gnomAD X-46853513-A-G, REVEL 0.31, CADD 20.20
- E48K (p.Glu48Lys), rs1242455423, ClinGen CA413038872, ClinVar RCV001352468, TOPMed rs1242455423, REVEL 0.33, CADD 22.60, Uncertain significance, not provided
- V50A (p.Val50Ala), gnomAD rs1556318536, REVEL 0.69, CADD 22.30
- V50L (p.Val50Leu), gnomAD X-46853521-G-C, REVEL 0.57, CADD 19.10
- G51V (p.Gly51Val), rs781992752, ExAC rs781992752, gnomAD rs781992752, REVEL 0.61, CADD 21.60, Variant assessed as somatic; moderate impact.
- G51D (p.Gly51Asp), gnomAD X-46853525-G-A, REVEL 0.82, CADD 25.60
- R52C (p.Arg52Cys), NCI-TCGA Cosmic COSV5446, TOPMed rs1924896260, REVEL 0.85, CADD 25.40, Variant assessed as somatic; moderate impact.
- R52H (p.Arg52His), rs782127844, ClinGen CA10394186, NCI-TCGA Cosmic COSV9950, ClinVar RCV002007758, REVEL 0.84, CADD 26.60, Uncertain significance, not provided
- R52S (p.Arg52Ser), gnomAD X-46853527-C-A, REVEL 0.88, CADD 24.60
- P54L (p.Pro54Leu), rs2519913794, ClinGen CA413038914, ClinVar RCV002979639, Uncertain significance, not provided
- P54P (p.Pro54Pro), rs782744976, gnomAD X-46853535-T-C, CADD 13.10
- G55R (p.Gly55Arg), rs1924896657, ClinGen CA413038915, ClinVar RCV001073339, ClinVar RCV001862802, AlphaMissense 0.40, MetaLR 0.91, Uncertain significance, not provided; Retinal dystrophy
- G55V (p.Gly55Val), rs2519913806, ClinGen CA413038920, ClinVar RCV002994046, Uncertain significance, not provided
- T56M (p.Thr56Met), rs1201646093, ClinGen CA413038926, NCI-TCGA Cosmic COSV5446, ClinVar RCV001211919, REVEL 0.28, AlphaMissense 0.07, Conflicting interpretations, not provided
- T56R (p.Thr56Arg), rs1201646093, ClinGen CA413038925, ClinVar RCV003863711, AlphaMissense 0.07, MetaLR 0.61, Uncertain significance, not provided
- T56A (p.Thr56Ala), gnomAD X-46853539-A-G, REVEL 0.24, CADD 18.90
- T56K (p.Thr56Lys), gnomAD X-46853540-C-A, REVEL 0.21, CADD 10.40
- T56T (p.Thr56Thr), rs371935908, gnomAD X-46853541-G-T, CADD 7.42
- V57A (p.Val57Ala), rs2519913839, ClinGen CA413038931, ClinVar RCV003027493, REVEL 0.49, CADD 23.50, Uncertain significance, not provided
- V57V (p.Val57Val), rs1924897055, gnomAD X-46853544-A-G, CADD 8.18
- A58P (p.Ala58Pro), gnomAD X-46853545-G-C, REVEL 0.45, CADD 21.70
- G59* (p.Gly59Ter), rs2147081178, ClinGen CA413038941, ClinVar RCV001863498, Ensembl rs2147081178, Pathogenic
- G59E (p.Gly59Glu), NCI-TCGA Cosmic COSV9950, Variant assessed as somatic; moderate impact.
- Q60* (p.Gln60Ter), rs1924897230, ClinGen CA413038946, ClinVar RCV001075521, Ensembl rs1924897230, Likely pathogenic
- I64T (p.Ile64Thr), rs782712704, ClinGen CA10394190, ClinVar RCV001340990, ExAC rs782712704, REVEL 0.95, CADD 25.40, Uncertain significance, not provided
- I64V (p.Ile64Val), TOPMed rs1924897310
Public RP2 analysis runs
- RP2 analysis run — RP2 (661 variants) — completed 2026-08-22