PMP22 (Peripheral myelin protein 22) variants and mutations
PMP22 (also known as Peripheral myelin protein 22) is a human protein-coding gene encoding a peripheral myelin protein 22 protein. Its dosage is critical for normal Schwann-cell myelin formation and stability in peripheral nerves. Duplication causes Charcot-Marie-Tooth disease type 1A, deletion causes hereditary neuropathy with liability to pressure palsies, and point variants cause additional neuropathies. This analysis covers 423 PMP22 variants and mutations. Of these, 85% have computational variant effect predictions. Disease context includes Charcot-Marie-Tooth disease type 1A, Dejerine-Sottas syndrome, and Charcot-Marie-Tooth disease type 1E. Example PMP22 variants include L3V, S7N, and I8M.
Variant analysis overview
- Gene: PMP22
- Protein: Peripheral myelin protein 22
- UniProt accession: Q01453
- Organism: Homo sapiens
- Variants analyzed: 423
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 261 unspecified-consequence records; 102 missense variants; 9 stop-gained variants; 24 synonymous variants; 14 frameshift variants; 1 in-frame deletions; 5 stop lost; 1 stop retained variant; 1 splice-region variants; 4 substitution
- Prediction scores: 359 variants have prediction scores (85% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Charcot-Marie-Tooth disease type 1A, Dejerine-Sottas syndrome, Charcot-Marie-Tooth disease type 1E, hereditary neuropathy with liability to pressure palsies, Charcot-Marie-Tooth disease type 3, Guillain-Barre syndrome, familial, Roussy-Lévy syndrome, Charcot-Marie-Tooth disease type 1, Charcot-Marie-Tooth disease, hereditary disease, Tip-toe gait, placental retention.
Protein structure and variant hotspots
- Protein features: 4 transmembrane segments; 1 post-translational modification sites.
- Structural context: 251 variants have structural context.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable PMP22 variants
Examples include L3V, S7N, I8M, I8N, I8S, I9N, I9V, L11R. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- L3V (p.Leu3Val), gnomAD rs1240600731, REVEL 0.31, CADD 21.60
- S7N (p.Ser7Asn), gnomAD rs1268254887, REVEL 0.28, CADD 22.80
- I8M (p.Ile8Met), cosmic curated COSV56603
- I8N (p.Ile8Asn), rs2508227523, ClinGen CA398271756, ClinVar RCV003742032, Uncertain significance, Charcot-Marie-Tooth disease, type I
- I8S (p.Ile8Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- I9N (p.Ile9Asn), rs2508227470, ClinGen CA398271751, ClinVar RCV002306066, REVEL 0.53, CADD 29.30, Uncertain significance, not provided
- I9V (p.Ile9Val), rs138515303, ClinGen CA8403455, ClinVar RCV001338852, ESP rs138515303, REVEL 0.23, CADD 22.20, Uncertain significance, Charcot-Marie-Tooth disease, type I
- L11R (p.Leu11Arg), rs1567719334, ClinGen CA398271736, ClinVar RCV000685969, Ensembl rs1567719334, AlphaMissense 0.97, MetaLR 0.74, Uncertain significance, Charcot-Marie-Tooth disease, type I
- L11V (p.Leu11Val), gnomAD rs1214377627, REVEL 0.34, CADD 24.70
- H12Q (p.His12Gln), rs104894622, ClinGen CA398271729, ClinVar RCV002900303, UniProt VAR 006359, REVEL 0.74, CADD 24.20, Pathogenic, Inborn genetic diseases; Charcot-Marie-Tooth disease, type I; not provided
- H12R (p.His12Arg), rs1909248652, ClinGen CA398271731, ClinVar RCV001036010, ClinVar RCV001548774, AlphaMissense 0.99, MetaLR 0.63, Pathogenic, not provided; Charcot-Marie-Tooth disease, type I
- H12Y (p.His12Tyr), rs2150710219, ClinGen CA398271733, ClinVar RCV002251247, Ensembl rs2150710219, REVEL 0.77, CADD 27.70, Likely pathogenic, Dejerine-Sottas disease
- V13A (p.Val13Ala), rs1909248074, ClinGen CA398271725, ClinVar RCV001239205, Ensembl rs1909248074, AlphaMissense 0.28, MetaLR 0.50, Uncertain significance, Charcot-Marie-Tooth disease, type I
- A14T (p.Ala14Thr), TOPMed rs1909247211, REVEL 0.29, CADD 22.20
- V15M (p.Val15Met), cosmic curated COSV10516, REVEL 0.44, CADD 25.00
- L16P (p.Leu16Pro), rs104894617, ClinGen CA340784, ClinVar RCV000008940, ClinVar RCV000685070, REVEL 0.80, CADD 32.00, Pathogenic, Charcot-Marie-Tooth disease, type I
- V17M (p.Val17Met), TOPMed rs929552332, REVEL 0.67, CADD 28.40
- L18R (p.Leu18Arg), rs1597635677, ClinGen CA398271697, ClinVar RCV000789514, Ensembl rs1597635677, AlphaMissense 0.98, MetaLR 0.75, Uncertain significance, Charcot-Marie-Tooth disease
- L18V (p.Leu18Val), cosmic curated COSV56601
- L19P (p.Leu19Pro), rs1597635666, ClinGen CA398271694, ClinVar RCV000789525, TOPMed rs1597635666, REVEL 0.92, CADD 32.00, Uncertain significance, Dejerine-Sottas disease
- L19Q (p.Leu19Gln), TOPMed rs1597635666, Uncertain significance, in DSS
- F20L (p.Phe20Leu), rs1436741083, ClinGen CA398271685, ClinVar RCV002360138, gnomAD rs1436741083, REVEL 0.40, CADD 22.90, Uncertain significance, Inborn genetic diseases
- V21L (p.Val21Leu), gnomAD rs1344381247, REVEL 0.52, CADD 23.60, Uncertain significance, Charcot-Marie-Tooth disease, type I; not provided
- S22F (p.Ser22Phe), rs104894625, ClinGen CA254390, ClinVar RCV000008958, ClinVar RCV000008959, REVEL 0.75, CADD 32.00, Pathogenic, Charcot-Marie-Tooth disease, type IA; Hereditary liability to pressure palsies
- S22P (p.Ser22Pro), rs1300756669, ClinGen CA398271676, ClinVar RCV003742526, AlphaMissense 0.61, MetaLR 0.47, Uncertain significance, Charcot-Marie-Tooth disease, type I
- S22T (p.Ser22Thr), gnomAD rs1300756669, REVEL 0.30, AlphaMissense 0.61
- S22Y (p.Ser22Tyr), rs104894625, ClinGen CA398271674, ClinVar RCV006436806, ClinVar RCV006556149, REVEL 0.73, CADD 32.00, Uncertain significance, not provided; Charcot-Marie-Tooth disease, type I
- T23K (p.Thr23Lys), rs906563423, ClinGen CA288109904, ClinVar RCV002039305, ClinVar RCV005409841, AlphaMissense 0.98, MetaLR 0.83, Pathogenic/Likely pathogenic, Charcot-Marie-Tooth disease, type IA; Charcot-Marie-Tooth disease, type I
- T23M (p.Thr23Met), rs906563423, ClinGen CA288109902, ClinVar RCV002995929, ClinVar RCV003989144, REVEL 0.80, AlphaMissense 0.98, Uncertain significance, Charcot-Marie-Tooth disease, type I; Charcot-Marie-Tooth disease, type IA
- T23R (p.Thr23Arg), rs906563423, ClinGen CA16615515, ClinVar RCV000471834, ClinVar RCV000789510, REVEL 0.85, AlphaMissense 0.98, Pathogenic/Likely pathogenic, not provided; Charcot-Marie-Tooth disease, type I; Charcot-Marie-Tooth disease
- I24M (p.Ile24Met), rs371373574, ClinGen CA398271663, ClinVar RCV001752044, ClinVar RCV003581799, AlphaMissense 0.22, MetaLR 0.69, Uncertain significance, Charcot-Marie-Tooth disease, type I; not provided
- I24V (p.Ile24Val), gnomAD rs1336298802, REVEL 0.41, CADD 23.10
- V25G (p.Val25Gly), rs765741053, ClinGen CA8403451, ClinVar RCV001123656, ClinVar RCV001123657, REVEL 0.61, CADD 26.20, Uncertain significance, Charcot-Marie-Tooth disease, type I; not provided; Hereditary liability to press
- V25I (p.Val25Ile), rs2508226786, ClinGen CA398271660, ClinVar RCV002285781, ClinVar RCV005096047, REVEL 0.50, CADD 24.80, Uncertain significance, Charcot-Marie-Tooth disease, type I; not provided
- W28* (p.Trp28Ter), rs1555568475, cosmic curated COSV10461, ClinGen CA398271192, ClinVar RCV000638157, Pathogenic, in CMT1E
- W28C (p.Trp28Cys), rs1442525908, ClinGen CA398271186, cosmic curated COSV56603, ClinVar RCV001027475, REVEL 0.87, CADD 29.00, Uncertain significance, Charcot-Marie-Tooth disease, type I
- W28R (p.Trp28Arg), rs104894626, ClinGen CA342724, ClinVar RCV000023072, ClinVar RCV002512924, AlphaMissense 1.00, MetaLR 0.96, Likely pathogenic, Charcot-Marie-Tooth disease, type I; not provided
- I29M (p.Ile29Met), 1000Genomes rs201192820, ExAC rs201192820, TOPMed rs201192820, gnomAD rs201192820, REVEL 0.17, CADD 13.40, Likely benign
- I29V (p.Ile29Val), Ensembl rs1909090808, REVEL 0.28, CADD 7.92
- V30L (p.Val30Leu), ESP rs377335295, ExAC rs377335295, TOPMed rs377335295, gnomAD rs377335295, REVEL 0.51, CADD 14.10, Likely benign, in HNPP
- V30M (p.Val30Met), rs377335295, ClinGen CA8403434, ClinVar RCV000790166, ClinVar RCV000796876, REVEL 0.65, CADD 19.40, Conflicting interpretations, Charcot-Marie-Tooth disease, type I; not provided
- G31D (p.Gly31Asp), gnomAD rs1451714453, REVEL 0.59, CADD 22.40
- G31S (p.Gly31Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- N32I (p.Asn32Ile), cosmic curated COSV10039
- N32S (p.Asn32Ser), ESP rs373322590, ExAC rs373322590, TOPMed rs373322590, gnomAD rs373322590, REVEL 0.14, CADD 15.40
- G33E (p.Gly33Glu), rs754175558, ClinGen CA8403431, ClinVar RCV001237650, ExAC rs754175558, REVEL 0.22, CADD 15.30, Uncertain significance, Charcot-Marie-Tooth disease, type I
- G33V (p.Gly33Val), cosmic curated COSV10039
- H34Q (p.His34Gln), rs779654897, ExAC rs779654897, TOPMed rs779654897, gnomAD rs779654897, REVEL 0.28, CADD 4.53, Uncertain significance, Charcot-Marie-Tooth disease, type IA
- H34Y (p.His34Tyr), rs756458019, ClinGen CA8403429, ClinVar RCV000638156, ClinVar RCV002438689, REVEL 0.20, CADD 14.70, Likely benign, Charcot-Marie-Tooth disease, type I; Inborn genetic diseases
- A35G (p.Ala35Gly), ExAC rs765235223, gnomAD rs765235223, REVEL 0.14, CADD 15.30, Uncertain significance, not provided
- A35P (p.Ala35Pro), ExAC rs750000952, TOPMed rs750000952, gnomAD rs750000952, REVEL 0.52, CADD 8.00, Uncertain significance
- A35T (p.Ala35Thr), rs750000952, ClinGen CA8403425, NCI-TCGA Cosmic COSV5660, cosmic curated COSV56601, REVEL 0.18, CADD 0.30, Conflicting interpretations, Charcot-Marie-Tooth disease, type I; not provided; Tip-toe gait
- A35V (p.Ala35Val), ExAC rs765235223, gnomAD rs765235223, REVEL 0.17, CADD 16.30
- T36A (p.Thr36Ala), rs2508212355, ClinGen CA398271080, ClinVar RCV002410920, Uncertain significance, Inborn genetic diseases
- D37H (p.Asp37His), rs1444447898, ClinGen CA398271064, ClinVar RCV003488290, gnomAD rs1444447898, AlphaMissense 0.70, MetaLR 0.76, Uncertain significance, not provided
- D37N (p.Asp37Asn), rs1444447898, ClinGen CA398271067, ClinVar RCV002833787, gnomAD rs1444447898, REVEL 0.54, AlphaMissense 0.70, Uncertain significance, Charcot-Marie-Tooth disease, type I
- D37V (p.Asp37Val), rs104894627, ClinGen CA119626, ClinVar RCV000008955, UniProt VAR 009660, AlphaMissense 0.98, MetaLR 0.84, Pathogenic, Charcot-Marie-Tooth disease, type 1a, with focally folded myelin sheaths
- L38I (p.Leu38Ile), Ensembl rs1053394734
- L38P (p.Leu38Pro), rs1234608261, ClinGen CA398271050, ClinVar RCV001904101, TOPMed rs1234608261, REVEL 0.95, CADD 29.40, Uncertain significance, Charcot-Marie-Tooth disease, type I
- W39* (p.Trp39Ter), rs797044846, ClinGen CA10604162, cosmic curated COSV10039, ClinVar RCV000297207, AlphaMissense 1.00, MetaLR 0.96, Pathogenic
- W39C (p.Trp39Cys), rs797044846, ClinGen CA347450, ClinVar RCV000195195, ClinVar RCV000790172, AlphaMissense 1.00, MetaLR 0.96, Uncertain significance, Charcot-Marie-Tooth disease
- Q40H (p.Gln40His), ExAC rs761801976, gnomAD rs761801976, REVEL 0.61, CADD 23.20
- C42R (p.Cys42Arg), rs2508212058, ClinGen CA398270963, ClinVar RCV003152871, ClinVar RCV003581894, Uncertain significance, Charcot-Marie-Tooth disease, type I; Charcot-Marie-Tooth disease, type IA; not p
- C42Y (p.Cys42Tyr), rs2508212037, ClinGen CA398270949, ClinVar RCV003741684, ClinVar RCV006562895, Uncertain significance, Charcot-Marie-Tooth disease, type I; not provided
- S43T (p.Ser43Thr), Ensembl rs539999617
- T44A (p.Thr44Ala), ExAC rs112651887, TOPMed rs112651887, gnomAD rs112651887, Uncertain significance
- T44S (p.Thr44Ser), rs112651887, ClinGen CA8403421, ClinVar RCV000688458, ExAC rs112651887, REVEL 0.19, CADD 13.30, Uncertain significance, Charcot-Marie-Tooth disease, type I
- S45F (p.Ser45Phe), rs1259742235, ClinGen CA398270896, cosmic curated COSV56602, ClinVar RCV001324390, REVEL 0.18, CADD 17.40, Uncertain significance, Charcot-Marie-Tooth disease, type I
- S45P (p.Ser45Pro), NCI-TCGA Cosmic COSV1003, cosmic curated COSV10039, Variant assessed as somatic; moderate impact.
- S46F (p.Ser46Phe), NCI-TCGA Cosmic COSV5660, cosmic curated COSV56602, REVEL 0.28, CADD 16.30, Variant assessed as somatic; moderate impact.
- S47* (p.Ser47Ter), cosmic curated COSV56603
- S47L (p.Ser47Leu), rs1213064078, NCI-TCGA Cosmic COSV5660, cosmic curated COSV56603, REVEL 0.17, CADD 17.50, Variant assessed as somatic; moderate impact.
- G48E (p.Gly48Glu), NCI-TCGA Cosmic COSV5660, cosmic curated COSV56602, Variant assessed as somatic; moderate impact.
- N49H (p.Asn49His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V50D (p.Val50Asp), TOPMed rs1446193946
- V50I (p.Val50Ile), cosmic curated COSV56603
- H51R (p.His51Arg), rs368908933, ClinGen CA337251, ClinVar RCV000762229, ClinVar RCV001087677, REVEL 0.21, CADD 14.80, Conflicting interpretations, Charcot-Marie-Tooth disease; Charcot-Marie-Tooth disease, type I; not provided
- H51Y (p.His51Tyr), gnomAD rs923608028, REVEL 0.22, CADD 15.40
- H52N (p.His52Asn), gnomAD rs1243991145, REVEL 0.28, CADD 20.60
- H52Y (p.His52Tyr), gnomAD 17-15239526-G-A, CADD 12.30
- F54V (p.Phe54Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S55P (p.Ser55Pro), NCI-TCGA Cosmic COSV5660, cosmic curated COSV56602, Variant assessed as somatic; moderate impact.
- S56L (p.Ser56Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S57* (p.Ser57Ter), rs1909079392, ClinGen CA398270684, ClinVar RCV001173913, Ensembl rs1909079392, CADD 39.00, Likely pathogenic
- S57L (p.Ser57Leu), cosmic curated COSV56603
- P58Q (p.Pro58Gln), rs745939923, ClinGen CA8403418, ClinVar RCV000688100, ClinVar RCV005702288, REVEL 0.09, CADD 9.67, Uncertain significance, Inborn genetic diseases; Charcot-Marie-Tooth disease, type I
- P58S (p.Pro58Ser), rs772242644, ClinGen CA8403419, ClinVar RCV001212797, ExAC rs772242644, REVEL 0.20, CADD 1.50, Uncertain significance, Charcot-Marie-Tooth disease, type I
- P58L (p.Pro58Leu), gnomAD 17-15239546-G-A, CADD 9.96
- P58T (p.Pro58Thr), gnomAD 17-15239580-G-T, CADD 9.57
- N59S (p.Asn59Ser), ExAC rs779004441, TOPMed rs779004441, gnomAD rs779004441, REVEL 0.17, CADD 16.50
- E60K (p.Glu60Lys), rs2508211197, ClinGen CA398270649, ClinVar RCV002404200, ClinVar RCV003581861, REVEL 0.66, CADD 34.00, Uncertain significance, Charcot-Marie-Tooth disease, type I; Charcot-Marie-Tooth disease, type IA; Inbor
- E60E (p.Glu60Glu), rs1223037928, gnomAD 17-15239610-T-C, CADD 15.20
- W61* (p.Trp61Ter), rs1597608203, ClinGen CA398268441, ClinVar RCV000789528, ClinVar RCV003581719, AlphaMissense 0.99, MetaLR 0.84, Pathogenic
- W61C (p.Trp61Cys), TOPMed rs1597608203, REVEL 0.81, AlphaMissense 0.99, Pathogenic
- W61L (p.Trp61Leu), cosmic curated COSV10039, REVEL 0.76, CADD 27.70
- L62P (p.Leu62Pro), ExAC rs756046682, TOPMed rs756046682, gnomAD rs756046682, Uncertain significance
- L62R (p.Leu62Arg), rs756046682, ClinGen CA334283, ClinVar RCV000168113, ClinVar RCV000765330, REVEL 0.93, CADD 29.50, Uncertain significance, not specified; Charcot-Marie-Tooth disease, type I; Guillain-Barre syndrome, fam
- Q63L (p.Gln63Leu), ExAC rs752712529, gnomAD rs752712529
- S64F (p.Ser64Phe), rs1311837830, ClinGen CA398268383, ClinVar RCV001909184, ClinVar RCV004042590, REVEL 0.78, CADD 29.40, Uncertain significance, Charcot-Marie-Tooth disease, type I; Inborn genetic diseases
- S64Y (p.Ser64Tyr), NCI-TCGA Cosmic COSV5660, cosmic curated COSV56603, Variant assessed as somatic; moderate impact.
- S64T (p.Ser64Thr), gnomAD 17-15239600-A-T, REVEL 0.41, CADD 23.30
- V65F (p.Val65Phe), rs1597608152, ClinGen CA398268368, ClinVar RCV000790157, Ensembl rs1597608152, AlphaMissense 0.97, MetaLR 0.88, Uncertain significance, Charcot-Marie-Tooth disease
- V65I (p.Val65Ile), rs779700333, gnomAD 17-15239544-C-T, CADD 10.60
- V65L (p.Val65Leu), rs769945527, gnomAD 17-15239550-C-G, CADD 9.35
- Q66P (p.Gln66Pro), rs1907131144, ClinGen CA398268346, ClinVar RCV001175246, Ensembl rs1907131144, AlphaMissense 0.98, MetaLR 0.87, Uncertain significance, Hereditary liability to pressure palsies
- A67P (p.Ala67Pro), rs104894623, ClinGen CA340786, ClinVar RCV000008951, ClinVar RCV000992662, AlphaMissense 0.99, MetaLR 0.88, Pathogenic/Likely pathogenic, Charcot-Marie-Tooth disease, type I; not provided
- A67S (p.Ala67Ser), TOPMed rs104894623, Pathogenic, in HNPP
- A67T (p.Ala67Thr), rs104894623, ClinGen CA254388, ClinVar RCV000008956, ClinVar RCV001173915, AlphaMissense 0.99, MetaLR 0.88, Conflicting interpretations, Charcot-Marie-Tooth disease, type I; Charcot-Marie-Tooth disease; not provided
- T68A (p.Thr68Ala), NCI-TCGA Cosmic COSV5660, cosmic curated COSV56602, Variant assessed as somatic; moderate impact.
- T68I (p.Thr68Ile), rs2150676849, ClinGen CA398268304, ClinVar RCV002034891, NCI-TCGA TCGA novel, AlphaMissense 0.44, MetaLR 0.65, Uncertain significance, Inborn genetic diseases; Charcot-Marie-Tooth disease, type I
- M69K (p.Met69Lys), rs104894620, ClinGen CA119618, ClinVar RCV000008947, ClinVar RCV000494533, AlphaMissense 0.98, MetaLR 0.87, Pathogenic, Charcot-Marie-Tooth disease, type I; not provided; Charcot-Marie-Tooth disease
- M69R (p.Met69Arg), rs104894620, ClinGen CA398268285, ClinVar RCV000790164, ClinVar RCV005092377, AlphaMissense 0.98, MetaLR 0.87, Likely pathogenic, Charcot-Marie-Tooth disease, type I
- M69T (p.Met69Thr), rs104894620, ClinGen CA288098399, ClinVar RCV000638164, ClinVar RCV001731826, AlphaMissense 0.98, MetaLR 0.87, Conflicting interpretations, not provided; Inborn genetic diseases; Charcot-Marie-Tooth disease, type I
- I70L (p.Ile70Leu), Ensembl rs1907129282, REVEL 0.79, CADD 25.00
- I70V (p.Ile70Val), gnomAD 17-15239582-T-C, REVEL 0.43, CADD 18.40
- L71P (p.Leu71Pro), rs940401899, ClinGen CA398268247, ClinVar RCV000790143, TOPMed rs940401899, AlphaMissense 0.99, MetaLR 0.87, Uncertain significance, Dejerine-Sottas disease
- L71Q (p.Leu71Gln), rs940401899, ClinGen CA288098392, ClinVar RCV003581256, ClinVar RCV005707174, REVEL 0.97, AlphaMissense 0.99, Uncertain significance, Inborn genetic diseases; Charcot-Marie-Tooth disease, type I
- S72* (p.Ser72Ter), rs104894621, ClinGen CA398268233, ClinVar RCV002000141, Ensembl rs104894621, AlphaMissense 1.00, MetaLR 0.89, Pathogenic, in DSS
- S72L (p.Ser72Leu), rs104894621, ClinGen CA119620, ClinVar RCV000008948, ClinVar RCV000456500, AlphaMissense 1.00, MetaLR 0.89, Pathogenic, PMP22-related disorder; Inborn genetic diseases; Charcot-Marie-Tooth disease, ty
- S72P (p.Ser72Pro), rs1597608086, ClinGen CA398268237, ClinVar RCV000789526, ClinVar RCV002535807, AlphaMissense 0.99, MetaLR 0.88, Pathogenic, Charcot-Marie-Tooth disease, type I
- S72W (p.Ser72Trp), rs104894621, ClinGen CA398268231, ClinVar RCV000790174, ClinVar RCV000802360, AlphaMissense 1.00, MetaLR 0.89, Pathogenic/Likely pathogenic, Charcot-Marie-Tooth disease, type I; not provided; Dejerine-Sottas disease
- I73N (p.Ile73Asn), rs1049906036, ClinGen CA288098387, ClinVar RCV001752664, TOPMed rs1049906036, REVEL 0.61, CADD 27.10, Uncertain significance, not provided
- I74M (p.Ile74Met), gnomAD 17-15239568-G-C, REVEL 0.79, CADD 24.70
- S76I (p.Ser76Ile), rs1597608049, ClinGen CA398268149, ClinVar RCV000790175, Ensembl rs1597608049, AlphaMissense 0.88, MetaLR 0.84, Uncertain significance, Dejerine-Sottas disease
- S76R (p.Ser76Arg), rs1555565283, ClinGen CA398268148, ClinVar RCV000517250, ClinVar RCV006463214, AlphaMissense 1.00, MetaLR 0.80, Conflicting interpretations, not provided; Charcot-Marie-Tooth disease, type I
- I77V (p.Ile77Val), rs936874481, ClinGen CA288098372, ClinVar RCV003871269, TOPMed rs936874481, REVEL 0.23, CADD 15.20, Uncertain significance, Charcot-Marie-Tooth disease, type I
- L78M (p.Leu78Met), ExAC rs766656618, gnomAD rs766656618, REVEL 0.41, CADD 23.80
- L78P (p.Leu78Pro), rs1555565276, ClinGen CA398268114, ClinVar RCV000498886, ClinVar RCV000518311, AlphaMissense 0.89, MetaLR 0.82, Conflicting interpretations, Charcot-Marie-Tooth disease, type I; not specified; not provided
- S79C (p.Ser79Cys), rs104894618, ClinGen CA254385, ClinVar RCV000008941, ClinVar RCV002512923, AlphaMissense 0.73, MetaLR 0.85, Pathogenic, Charcot-Marie-Tooth disease, type I
- S79F (p.Ser79Phe), rs104894618, ClinGen CA398268094, ClinVar RCV001385499, Ensembl rs104894618, AlphaMissense 0.73, MetaLR 0.85, Pathogenic, Charcot-Marie-Tooth disease, type I
- S79P (p.Ser79Pro), rs863225027, ClinGen CA398268103, ClinVar RCV000790146, ClinVar RCV003581730, AlphaMissense 0.97, MetaLR 0.79, Pathogenic, Charcot-Marie-Tooth disease, type I
- S79T (p.Ser79Thr), rs863225027, ClinGen CA279110, ClinVar RCV000201185, ClinVar RCV001206556, AlphaMissense 0.97, MetaLR 0.79, Likely pathogenic, Charcot-Marie-Tooth disease, type IA; Charcot-Marie-Tooth disease, type I
- L80P (p.Leu80Pro), rs1597607967, ClinGen CA398268077, ClinVar RCV000790176, Ensembl rs1597607967, AlphaMissense 0.98, MetaLR 0.85, Uncertain significance, Dejerine-Sottas disease
- L80R (p.Leu80Arg), rs1597607967, ClinGen CA398268079, ClinVar RCV000790155, Ensembl rs1597607967, AlphaMissense 0.98, MetaLR 0.85, Uncertain significance, Dejerine-Sottas disease
- L80V (p.Leu80Val), rs773201903, ClinGen CA8403379, ClinVar RCV002459555, ExAC rs773201903, REVEL 0.69, CADD 23.40, Uncertain significance, Inborn genetic diseases
- F81L (p.Phe81Leu), rs748551014, ClinGen CA8403377, ClinVar RCV002015256, ExAC rs748551014, REVEL 0.55, CADD 23.10, Uncertain significance, Charcot-Marie-Tooth disease, type I
- L82P (p.Leu82Pro), rs878853113, ClinGen CA10581428, ClinVar RCV000224582, ClinVar RCV001050263, AlphaMissense 0.94, MetaLR 0.80, Conflicting interpretations, Charcot-Marie-Tooth disease, type I; not provided
- L82F (p.Leu82Phe), rs925414870, gnomAD 17-15239529-G-A, CADD 10.10
- F83L (p.Phe83Leu), cosmic curated COSV56601, Ensembl rs1429141312, NCI-TCGA Cosmic COSV5660, cosmic curated COSV56603, REVEL 0.80, CADD 27.20, Variant assessed as somatic; moderate impact.
- F84F (p.Phe84Phe), gnomAD 17-15239538-G-A, CADD 12.60
- C85* (p.Cys85Ter), rs755701957, ClinGen CA398267979, ClinVar RCV001173914, TOPMed rs755701957, AlphaMissense 0.68, MetaLR 0.76, Likely pathogenic
- C85W (p.Cys85Trp), rs755701957, ClinGen CA288098333, ClinVar RCV000638175, ClinVar RCV000857020, REVEL 0.59, AlphaMissense 0.68, Uncertain significance, Inborn genetic diseases; Hereditary liability to pressure palsies; Guillain-Barr
- Q86* (p.Gln86Ter), rs11545341, ClinGen CA398267972, ClinVar RCV000789532, ClinVar RCV000992663, AlphaMissense 0.94, MetaLR 0.87, Pathogenic
- Q86K (p.Gln86Lys), Ensembl rs11545341, Pathogenic
- L87I (p.Leu87Ile), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L87P (p.Leu87Pro), rs1907114176, ClinGen CA398267949, ClinVar RCV001093239, ClinVar RCV004546600, AlphaMissense 0.99, MetaLR 0.87, Uncertain significance, not provided; Dejerine-Sottas disease; Roussy-Lévy syndrome
- L87V (p.Leu87Val), gnomAD 17-15239531-G-C, REVEL 0.87, CADD 26.90
- F88L (p.Phe88Leu), TOPMed rs1907112676
- F88S (p.Phe88Ser), gnomAD 17-15239527-A-G, REVEL 0.88, CADD 30.00
- T89I (p.Thr89Ile), 1000Genomes rs189205303, TOPMed rs189205303, Uncertain significance
- T89N (p.Thr89Asn), rs189205303, ClinGen CA288098306, ClinVar RCV001122568, ClinVar RCV001122569, REVEL 0.52, CADD 23.80, Uncertain significance, Charcot-Marie-Tooth disease, type I; Hereditary liability to pressure palsies
- L90V (p.Leu90Val), rs147114400, ClinGen CA8403375, ClinVar RCV000796170, ClinVar RCV002424823, REVEL 0.62, CADD 23.30, Benign/Likely benign, Inborn genetic diseases; Charcot-Marie-Tooth disease, type I; not specified
- T91A (p.Thr91Ala), Ensembl rs1567704762, REVEL 0.19, CADD 22.20
- K92E (p.Lys92Glu), cosmic curated COSV56602, REVEL 0.76, CADD 27.50
- K92M (p.Lys92Met), TOPMed rs112232836, gnomAD rs112232836
- K92N (p.Lys92Asn), Ensembl rs1597607841
- K92R (p.Lys92Arg), cosmic curated COSV56602, TOPMed rs112232836, gnomAD rs112232836, REVEL 0.67, CADD 24.60
- K92K (p.Lys92Lys), gnomAD 17-15239439-C-T, CADD 0.78
- G93A (p.Gly93Ala), rs757021177, ClinGen CA8403372, ClinVar RCV002994167, ClinVar RCV003493974, REVEL 0.87, CADD 25.50, Uncertain significance, not specified; Charcot-Marie-Tooth disease, type I
- G93R (p.Gly93Arg), rs778693173, ExAC rs778693173, TOPMed rs778693173, gnomAD rs778693173, REVEL 0.92, CADD 27.10, Uncertain significance, Charcot-Marie-Tooth disease, type I; not provided
- G93V (p.Gly93Val), ExAC rs757021177, TOPMed rs757021177, gnomAD rs757021177, REVEL 0.91, CADD 27.10, Uncertain significance, in CMT1A
- G93W (p.Gly93Trp), rs778693173, ClinGen CA398267492, ClinVar RCV003741384, ExAC rs778693173, REVEL 0.92, CADD 28.90, Uncertain significance, Charcot-Marie-Tooth disease, type I
- G93E (p.Gly93Glu), gnomAD 17-15239512-C-T, REVEL 0.90, CADD 26.20
- G94D (p.Gly94Asp), gnomAD rs1305424913, REVEL 0.65, CADD 23.80
- G94S (p.Gly94Ser), rs1335714957, ClinGen CA398267486, cosmic curated COSV56602, ClinVar RCV003233171, REVEL 0.62, CADD 24.50, Uncertain significance, not provided; Charcot-Marie-Tooth disease, type I
- G94V (p.Gly94Val), gnomAD rs1305424913, REVEL 0.83, CADD 25.60
- G94fsX222, rs80338763, Conflicting interpretations
- G94SfsX16, rs864622678, Pathogenic
- R95K (p.Arg95Lys), rs1555565234, ClinGen CA398267475, ClinVar RCV000516786, ClinVar RCV001173923, REVEL 0.68, CADD 23.40, Uncertain significance, not specified; Charcot-Marie-Tooth disease
- R95C (p.Arg95Cys), rs863225028, gnomAD 17-15231073-G-A, CADD 0.79
- F96L (p.Phe96Leu), cosmic curated COSV10039, REVEL 0.89, CADD 29.20
- Y97L (p.Tyr97Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- Y97C (p.Tyr97Cys), gnomAD 17-15239500-T-C, REVEL 0.72, CADD 28.80
- I98L (p.Ile98Leu), ExAC rs748778392, gnomAD rs748778392, REVEL 0.20, CADD 15.90, Uncertain significance
- I98V (p.Ile98Val), rs748778392, ClinGen CA288098219, ClinVar RCV002027192, ExAC rs748778392, REVEL 0.23, CADD 18.20, Uncertain significance, Charcot-Marie-Tooth disease, type I
- T99I (p.Thr99Ile), rs1467889270, ClinGen CA398267441, ClinVar RCV003012182, gnomAD rs1467889270, REVEL 0.93, CADD 28.30, Uncertain significance, Charcot-Marie-Tooth disease, type I
- T99P (p.Thr99Pro), ExAC rs777109239, TOPMed rs777109239, gnomAD rs777109239, REVEL 0.95, CADD 28.90
- T99S (p.Thr99Ser), gnomAD 17-15239494-G-C, REVEL 0.70, CADD 26.80
- T99A (p.Thr99Ala), gnomAD 17-15239495-T-C, REVEL 0.88, CADD 27.40
- G100E (p.Gly100Glu), rs1597607638, ClinGen CA398267432, ClinVar RCV000789516, Ensembl rs1597607638, AlphaMissense 1.00, MetaLR 0.92, Uncertain significance, Dejerine-Sottas disease
Public PMP22 analysis runs
- PMP22 analysis run — PMP22 (423 variants) — completed 2026-08-19