PKP2 (Plakophilin-2) variants and mutations
PKP2 (also known as Plakophilin-2) is a human protein-coding gene encoding a plakophilin-2 protein. It organizes cardiac desmosomes and helps maintain both mechanical adhesion and electrical coupling between cardiomyocytes. Pathogenic variants are a major cause of arrhythmogenic cardiomyopathy and increase susceptibility to ventricular arrhythmias and sudden cardiac death. This analysis covers 762 PKP2 variants and mutations. Of these, 75% have computational variant effect predictions. Disease context includes Arrhythmogenic right ventricular dysplasia, arrhythmogenic right ventricular cardiomyopathy, and cardiomyopathy. Example PKP2 variants include M1L, M1T, and M1V.
Variant analysis overview
- Gene: PKP2
- Protein: Plakophilin-2
- UniProt accession: Q99959
- Organism: Homo sapiens
- Variants analyzed: 762
- Variant scope: all variants
- Completed: 2026-08-10
Variant and mutation evidence
- Variant composition: 499 unspecified-consequence records; 1 stop lost; 55 synonymous variants; 176 missense variants; 8 stop-gained variants; 15 frameshift variants; 2 splice-region variants; 3 in-frame deletions; 2 in-frame insertions; 1 substitution
- Prediction scores: 570 variants have prediction scores (75% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Arrhythmogenic right ventricular dysplasia, arrhythmogenic right ventricular cardiomyopathy, cardiomyopathy, Abnormality of the cardiovascular system, familial isolated arrhythmogenic right ventricular dysplasia, atrial fibrillation, cardiac arrhythmia, left ventricular noncompaction, ventricular tachycardia, hypertrophic cardiomyopathy, inherited retinal dystrophy, familial isolated arrhythmogenic ventricular dysplasia, left dominant form.
Protein structure and variant hotspots
- Protein features: 16 post-translational modification sites.
- PTM context: 11 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable PKP2 variants
Examples include M1L, M1T, M1V, A3S, P4T, G5A, G11S, Y12C. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1L (p.Met1Leu), rs794729107, ClinGen CA384371856, ClinVar RCV003508864, ClinGen CA384371855, MetaLR 0.30, MetaSVM -0.63, Likely pathogenic, Arrhythmogenic right ventricular dysplasia 9
- M1T (p.Met1Thr), rs1957129506, ClinGen CA384371851, ClinVar RCV001178978, ClinVar RCV001875915, MetaLR 0.35, MetaSVM -0.35, Likely pathogenic, Arrhythmogenic right ventricular cardiomyopathy; Cardiomyopathy; Arrhythmogenic
- M1V (p.Met1Val), rs794729107, ClinGen CA011630, ClinVar RCV002890496, ClinVar RCV006342608, MetaLR 0.30, MetaSVM -0.63, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; Cardiovascular phenotype; not prov
- A3S (p.Ala3Ser), rs2541385290, ClinGen CA384371825, ClinVar RCV003482057, REVEL 0.13, MetaLR 0.28, Uncertain significance, not provided
- P4T (p.Pro4Thr), rs1425675043, ClinGen CA384371818, ClinVar RCV003507743, REVEL 0.10, MetaLR 0.25, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- G5A (p.Gly5Ala), rs2541385249, ClinGen CA604480711, ClinVar RCV004018334, Likely pathogenic
- G11S (p.Gly11Ser), rs1250140346, ClinGen CA384371728, ClinVar RCV003532792, REVEL 0.47, MetaLR 0.65, Uncertain significance, Cardiomyopathy
- Y12C (p.Tyr12Cys), rs763433296, ClinGen CA037040, ClinVar RCV001178390, ClinVar RCV001352524, REVEL 0.70, MetaLR 0.66, Uncertain significance, Cardiovascular phenotype; Arrhythmogenic right ventricular cardiomyopathy; Cardi
- I13L (p.Ile13Leu), rs2541385099, ClinGen CA384371705, ClinVar RCV004014263, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- Q19E (p.Gln19Glu), rs1261917007, ClinGen CA384371634, ClinVar RCV004013215, REVEL 0.20, MetaLR 0.26, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- G23* (p.Gly23Ter), rs770498155, ClinGen CA384371581, ClinVar RCV003508117, CADD 36.00, Pathogenic
- D26N (p.Asp26Asn), rs143004808, ClinGen CA010689, cosmic curated COSV10608, ClinVar RCV000038225, REVEL 0.43, MetaLR 0.45, Benign/Likely benign, Hypertrophic cardiomyopathy; Cardiomyopathy; Cardiovascular phenotype
- S28Y (p.Ser28Tyr), NCI-TCGA TCGA novel, REVEL 0.57, MetaLR 0.59, Variant assessed as somatic; moderate impact.
- L30R (p.Leu30Arg), rs1957128191, ClinGen CA384371480, ClinVar RCV004016865, AlphaMissense 0.98, MetaLR 0.70, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- L32M (p.Leu32Met), rs2541384760, ClinGen CA384371469, ClinVar RCV003508174, REVEL 0.28, MetaLR 0.66, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- E35K (p.Glu35Lys), rs754791731, ClinGen CA026929, ClinVar RCV003532791, ClinVar RCV005692618, REVEL 0.38, MetaLR 0.54, Uncertain significance, Cardiomyopathy; Cardiovascular phenotype
- E35R (p.Glu35Arg), rs2541384720, ClinGen CA2582342495, ClinVar RCV003340737, Likely pathogenic
- A36V (p.Ala36Val), rs2541384684, ClinGen CA384371370, ClinVar RCV003120481, ClinVar RCV003618048, REVEL 0.24, MetaLR 0.42, Uncertain significance, not provided; Arrhythmogenic right ventricular dysplasia 9
- A41R (p.Ala41Arg), rs2541384623, ClinGen CA2580085401, ClinVar RCV003000162, Pathogenic
- G42E (p.Gly42Glu), rs2541384586, ClinGen CA384371241, ClinVar RCV003837804, ClinVar RCV004006107, REVEL 0.44, MetaLR 0.56, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; Arrhythmogenic right ventricular c
- S44P (p.Ser44Pro), rs2541384544, ClinGen CA2580085400, ClinVar RCV002380825, ClinVar RCV003618000, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; Cardiovascular phenotype
- G45D (p.Gly45Asp), rs2541384526, ClinGen CA384371190, ClinVar RCV003532790, REVEL 0.11, MetaLR 0.29, Uncertain significance, Cardiomyopathy
- R46A (p.Arg46Ala), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- R46P (p.Arg46Pro), NCI-TCGA Cosmic COSV5074, cosmic curated COSV50747, Variant assessed as somatic; moderate impact.
- G47R (p.Gly47Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- G48D (p.Gly48Asp), rs2541384477, ClinGen CA384371140, ClinVar RCV004015279, REVEL 0.17, MetaLR 0.19, Uncertain significance, Cardiomyopathy
- T50R (p.Thr50Arg), rs1402887591, ClinGen CA384371082, ClinVar RCV004015659, AlphaMissense 0.17, MetaLR 0.21, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- V51D (p.Val51Asp), rs397516997, ClinGen CA2697559159, ClinVar RCV003507167, Pathogenic
- R55W (p.Arg55Trp), rs2541384358, ClinGen CA384370962, ClinVar RCV003071783, REVEL 0.65, MetaLR 0.68, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- E58* (p.Glu58Ter), rs1197820814, ClinGen CA384370911, ClinVar RCV003317864, CADD 39.00, Pathogenic
- E58D (p.Glu58Asp), rs146708884, ClinGen CA011366, ClinVar RCV000038182, ClinVar RCV000250199, REVEL 0.17, MetaLR 0.22, Benign/Likely benign, Cardiovascular phenotype; not specified; not provided
- Q59A (p.Gln59Ala), rs2541384294, ClinGen CA2580085397, ClinVar RCV003025803, Pathogenic, in ARVD9
- Q59L (p.Gln59Leu), rs730880179, ClinGen CA384370877, ClinVar RCV002401789, ClinVar RCV003533235, REVEL 0.80, MetaLR 0.51, Conflicting interpretations, Arrhythmogenic right ventricular cardiomyopathy; Arrhythmogenic right ventricula
- Q62K (p.Gln62Lys), rs199601548, ClinGen CA010651, ClinVar RCV000148732, ClinVar RCV000183769, REVEL 0.44, MetaLR 0.28, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- A65T (p.Ala65Thr), rs143323961, ClinGen CA384370680, ClinVar RCV004015951, REVEL 0.31, MetaLR 0.56, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- K67Q (p.Lys67Gln), rs1555149950, ClinGen CA384370597, ClinVar RCV003508130, AlphaMissense 0.70, MetaLR 0.29, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- S70I (p.Ser70Ile), rs75909145, ClinGen CA011711, ClinVar RCV000038197, ClinVar RCV000206028, REVEL 0.15, MetaLR 0.19, Benign/Likely benign, Cardiovascular phenotype; not specified; not provided
- G75* (p.Gly75Ter), rs765852160, ClinGen CA384370368, ClinVar RCV003150764, CADD 52.00, SIFT 0.00, Likely pathogenic
- G75E (p.Gly75Glu), rs267603443, ClinGen CA235267475, NCI-TCGA Cosmic COSV5073, cosmic curated COSV50731, REVEL 0.46, MetaLR 0.79, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; not specified; Cardiomyopathy
- G75V (p.Gly75Val), NCI-TCGA Cosmic COSV5073, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, TOPMed rs267603443, Uncertain significance, Cardiovascular phenotype
- N76H (p.Asn76His), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, Variant assessed as somatic; moderate impact.
- N76S (p.Asn76Ser), rs1201224837, UniProt VAR 070276, Ensembl rs1201224837, REVEL 0.12, MetaLR 0.19
- L77F (p.Leu77Phe), NCI-TCGA Cosmic COSV5075, cosmic curated COSV50754, Variant assessed as somatic; moderate impact.
- L77I (p.Leu77Ile), NCI-TCGA Cosmic COSV5075, REVEL 0.36, MetaLR 0.65, Variant assessed as somatic; moderate impact.
- S82R (p.Ser82Arg), rs2541345132, ClinGen CA384366652, ClinVar RCV003487252, Uncertain significance, Cardiomyopathy
- P84S (p.Pro84Ser), rs756468173, ClinGen CA035712, NCI-TCGA Cosmic COSV5074, cosmic curated COSV50742, REVEL 0.56, MetaLR 0.85, Uncertain significance, Cardiovascular phenotype; not provided; Cardiomyopathy
- E85D (p.Glu85Asp), rs1366955346, NCI-TCGA Cosmic COSV5072, cosmic curated COSV50728, gnomAD rs1366955346, REVEL 0.41, MetaLR 0.69, Likely benign
- E85Q (p.Glu85Gln), rs2137953226, ClinGen CA384366633, ClinVar RCV003171725, AlphaMissense 0.75, MetaLR 0.76, Uncertain significance, Cardiovascular phenotype
- E94K (p.Glu94Lys), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, Variant assessed as somatic; moderate impact.
- D96N (p.Asp96Asn), NCI-TCGA Cosmic COSV5073, cosmic curated COSV50739, MetaLR 0.30, MetaSVM -0.73, Variant assessed as somatic; moderate impact.
- D96Y (p.Asp96Tyr), rs2541344774, ClinGen CA384366555, ClinVar RCV004014109, ClinVar RCV006483826, REVEL 0.56, MetaLR 0.65, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; Arrhythmogenic right ventricular c
- G99V (p.Gly99Val), NCI-TCGA TCGA novel, MetaLR 0.29, MetaSVM -0.91, Variant assessed as somatic; moderate impact.
- R101C (p.Arg101Cys), rs796827562, ClinGen CA235267357, NCI-TCGA Cosmic COSV5073, cosmic curated COSV50730, REVEL 0.36, MetaLR 0.39, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy; Cardiomyopathy; Arrhythmogenic
- R101H (p.Arg101His), rs149542398, ClinGen CA012247, cosmic curated COSV50748, ClinVar RCV000038217, REVEL 0.19, MetaLR 0.33, Conflicting interpretations, Cardiovascular phenotype; not specified; Cardiomyopathy
- R101L (p.Arg101Leu), rs149542398, ClinGen CA235267349, ClinVar RCV002435993, ClinVar RCV003111558, REVEL 0.21, MetaLR 0.31, Uncertain significance, Cardiovascular phenotype; Arrhythmogenic right ventricular cardiomyopathy; Cardi
- P103L (p.Pro103Leu), NCI-TCGA Cosmic COSV5075, cosmic curated COSV50754, Ensembl rs1956960849, MetaLR 0.30, MetaSVM -0.72, Variant assessed as somatic; moderate impact.
- P103R (p.Pro103Arg), rs1956960817, ClinGen CA1139768740, ClinVar RCV003048230, REVEL 0.30, MetaLR 0.50, Pathogenic
- V104C (p.Val104Cys), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- D109A (p.Asp109Ala), rs756446946, ClinGen CA384366364, ClinVar RCV004015534, AlphaMissense 0.30, MetaLR 0.60, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- D109Y (p.Asp109Tyr), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, REVEL 0.48, MetaLR 0.58, Variant assessed as somatic; moderate impact.
- M110V (p.Met110Val), rs2541344445, ClinGen CA384366356, ClinVar RCV003533823, ClinVar RCV004287268, REVEL 0.10, MetaLR 0.24, Uncertain significance, Cardiomyopathy; Cardiovascular phenotype
- K112N (p.Lys112Asn), UniProt VAR 070277, REVEL 0.28, MetaLR 0.52
- A113S (p.Ala113Ser), rs1013290479, ClinGen CA384365516, ClinVar RCV002790263, ClinVar RCV004654028, REVEL 0.07, MetaLR 0.24, Uncertain significance, Cardiovascular phenotype; Arrhythmogenic right ventricular dysplasia 9
- T115A (p.Thr115Ala), rs2541343191, ClinGen CA384365505, ClinVar RCV002843518, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- E120K (p.Glu120Lys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R122C (p.Arg122Cys), rs759377911, ClinGen CA037071, NCI-TCGA Cosmic COSV5075, cosmic curated COSV50752, REVEL 0.25, MetaLR 0.39, Uncertain significance, Cardiovascular phenotype; Cardiomyopathy; Arrhythmogenic right ventricular dyspl
- W123* (p.Trp123Ter), rs760576804, ClinGen CA012280, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, CADD 36.00, SIFT 0.02, Pathogenic
- T127R (p.Thr127Arg), rs2541342943, ClinGen CA384365430, ClinVar RCV004016770, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- Q129L (p.Gln129Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- Q129S (p.Gln129Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- Y130C (p.Tyr130Cys), NCI-TCGA TCGA novel, REVEL 0.40, MetaLR 0.71, Variant assessed as somatic; moderate impact.
- Y130H (p.Tyr130His), rs2541342895, ClinGen CA384365413, ClinVar RCV003532786, Uncertain significance, Cardiomyopathy
- S132F (p.Ser132Phe), rs765241754, ClinGen CA384365395, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, AlphaMissense 0.19, MetaLR 0.63, Uncertain significance, Cardiomyopathy; Arrhythmogenic right ventricular cardiomyopathy
- K134Q (p.Lys134Gln), rs2541342733, ClinGen CA384365387, ClinVar RCV004013508, REVEL 0.29, MetaLR 0.60, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- E137A (p.Glu137Ala), rs2541342621, ClinGen CA384365366, ClinVar RCV004519049, Uncertain significance, Cardiovascular phenotype
- E137K (p.Glu137Lys), rs781739949, ClinGen CA037294, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, REVEL 0.29, MetaLR 0.60, Uncertain significance, not specified; not provided; Cardiomyopathy
- E138K (p.Glu138Lys), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, TOPMed rs1591829022, Variant assessed as somatic; moderate impact.
- S140F (p.Ser140Phe), rs150821281, ClinGen CA010672, ClinVar RCV000038218, ClinVar RCV000148729, REVEL 0.47, MetaLR 0.30, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- L141M (p.Leu141Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R142S (p.Arg142Ser), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, Variant assessed as somatic; moderate impact.
- R142K (p.Arg142Lys), NCI-TCGA Cosmic COSV5073, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, Variant assessed as somatic; moderate impact.
- R142M (p.Arg142Met), NCI-TCGA Cosmic COSV5073, cosmic curated COSV50736, NCI-TCGA Cosmic COSV9929, Variant assessed as somatic; moderate impact.
- H143Y (p.His143Tyr), rs2541342464, ClinGen CA384365321, ClinVar RCV003508863, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- P144S (p.Pro144Ser), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, MetaLR 0.83, MetaSVM 0.80, Variant assessed as somatic; moderate impact.
- L145R (p.Leu145Arg), rs1248218497, ClinGen CA384365279, ClinVar RCV004013740, AlphaMissense 0.48, MetaLR 0.67, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- L145V (p.Leu145Val), rs2541342424, ClinGen CA384365289, ClinVar RCV003002918, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- R146K (p.Arg146Lys), rs2541342360, ClinGen CA384365268, ClinVar RCV004008158, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- R147* (p.Arg147Ter), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, CADD 36.00, Variant assessed as somatic; high impact.
- E149D (p.Glu149Asp), rs778151977, ClinGen CA384365227, ClinVar RCV004013593, AlphaMissense 0.81, MetaLR 0.38, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- S155G (p.Ser155Gly), rs2541342135, ClinGen CA384365146, ClinVar RCV003486203, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- P156T (p.Pro156Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- E157Q (p.Glu157Gln), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, MetaLR 0.40, MetaSVM -0.74, Variant assessed as somatic; moderate impact.
- R158K (p.Arg158Lys), rs397517027, ClinGen CA012348, NCI-TCGA Cosmic COSV5072, cosmic curated COSV50725, REVEL 0.46, MetaLR 0.34, Conflicting interpretations, Cardiovascular phenotype; not specified; Cardiomyopathy
- H160Y (p.His160Tyr), rs1360804472, ClinGen CA384365071, NCI-TCGA Cosmic COSV5073, cosmic curated COSV50739, REVEL 0.18, MetaLR 0.25, Uncertain significance, Cardiomyopathy
- Y161C (p.Tyr161Cys), rs775789180, ClinGen CA037575, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, AlphaMissense 0.11, MetaLR 0.67, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- T162M (p.Thr162Met), rs759687672, ClinGen CA037611, ClinVar RCV001181600, ClinVar RCV001220028, REVEL 0.13, MetaLR 0.26, Uncertain significance, Cardiovascular phenotype; Arrhythmogenic right ventricular cardiomyopathy; Cardi
- H163Q (p.His163Gln), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H163R (p.His163Arg), rs2541341821, ClinGen CA384365020, ClinVar RCV003618575, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- S164N (p.Ser164Asn), rs2541341802, ClinGen CA384364991, ClinVar RCV003532785, Uncertain significance, Cardiomyopathy
- Y168C (p.Tyr168Cys), NCI-TCGA TCGA novel, MetaLR 0.56, MetaSVM -0.46, Variant assessed as somatic; moderate impact.
- S169G (p.Ser169Gly), rs139139859, ClinGen CA010682, ClinVar RCV000038222, ClinVar RCV000148728, REVEL 0.52, MetaLR 0.25, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- R171K (p.Arg171Lys), rs2541341631, ClinGen CA384364813, ClinVar RCV004013897, REVEL 0.15, MetaLR 0.30, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- Q173H (p.Gln173His), rs1387606757, ClinGen CA384364766, ClinVar RCV004016432, ClinVar RCV006348008, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy; Cardiovascular phenotype
- A174S (p.Ala174Ser), rs2137949857, ClinGen CA384364754, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, AlphaMissense 0.08, MetaLR 0.33, Uncertain significance, Cardiomyopathy
- H180R (p.His180Arg), rs2541341475, ClinGen CA384364632, ClinVar RCV002511481, ClinVar RCV006553348, REVEL 0.26, MetaLR 0.29, Uncertain significance, not provided; Arrhythmogenic right ventricular dysplasia 9; Cardiomyopathy
- E182K (p.Glu182Lys), NCI-TCGA TCGA novel, REVEL 0.25, MetaLR 0.42, Variant assessed as somatic; moderate impact.
- R185W (p.Arg185Trp), rs571569344, ClinGen CA037878, NCI-TCGA Cosmic COSV5072, cosmic curated COSV50726, REVEL 0.57, MetaLR 0.64, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; Arrhythmogenic right ventricular c
- A186V (p.Ala186Val), NCI-TCGA TCGA novel, REVEL 0.23, MetaLR 0.28, Variant assessed as somatic; moderate impact.
- A187T (p.Ala187Thr), rs200095747, ClinGen CA037962, NCI-TCGA Cosmic COSV5074, cosmic curated COSV50742, REVEL 0.13, MetaLR 0.15, Conflicting interpretations, not specified; Cardiovascular phenotype; Cardiomyopathy
- P192S (p.Pro192Ser), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, MetaLR 0.70, MetaSVM -0.38, Variant assessed as somatic; moderate impact.
- R193T (p.Arg193Thr), rs2541341255, ClinGen CA384364294, ClinVar RCV004014433, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- Y194C (p.Tyr194Cys), rs2541341229, ClinGen CA384364271, ClinVar RCV004160394, Uncertain significance, Cardiovascular phenotype
- A195V (p.Ala195Val), rs1041783952, ClinGen CA235266494, cosmic curated COSV50730, ClinVar RCV001184276, REVEL 0.44, MetaLR 0.64, Uncertain significance, Cardiomyopathy; Arrhythmogenic right ventricular dysplasia 9
- R196C (p.Arg196Cys), rs748957791, ClinGen CA012402, NCI-TCGA Cosmic COSV5073, cosmic curated COSV50735, REVEL 0.60, MetaLR 0.75, Uncertain significance, Cardiovascular phenotype; Arrhythmogenic right ventricular cardiomyopathy; Cardi
- I199N (p.Ile199Asn), rs2541341170, ClinGen CA384364139, ClinVar RCV003856065, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- V202I (p.Val202Ile), NCI-TCGA TCGA novel, REVEL 0.14, MetaLR 0.21, Variant assessed as somatic; moderate impact.
- S203C (p.Ser203Cys), rs2541341038, ClinGen CA384364079, ClinVar RCV004015133, ClinVar RCV006551090, Uncertain significance, Cardiomyopathy; Arrhythmogenic right ventricular cardiomyopathy
- R204H (p.Arg204His), rs755215178, ClinGen CA012412, NCI-TCGA Cosmic COSV5074, NCI-TCGA Cosmic COSV9929, REVEL 0.18, MetaLR 0.19, Conflicting interpretations, not specified; Cardiomyopathy; Cardiovascular phenotype
- R204L (p.Arg204Leu), NCI-TCGA Cosmic COSV5074, cosmic curated COSV50742, NCI-TCGA Cosmic COSV9929, REVEL 0.19, MetaLR 0.23, Variant assessed as somatic; moderate impact.
- A205P (p.Ala205Pro), rs2541340967, ClinGen CA384364031, ClinVar RCV002360380, Uncertain significance, Cardiovascular phenotype
- A205T (p.Ala205Thr), rs2541340967, ClinGen CA384364039, ClinVar RCV002632504, ClinVar RCV004009467, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; Arrhythmogenic right ventricular c
- R212H (p.Arg212His), rs1369618463, ClinGen CA384363873, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, REVEL 0.23, MetaLR 0.42, Conflicting interpretations, Arrhythmogenic right ventricular cardiomyopathy; not provided; Cardiomyopathy
- H213Y (p.His213Tyr), NCI-TCGA Cosmic COSV5073, cosmic curated COSV50730, Variant assessed as somatic; moderate impact.
- Y217* (p.Tyr217Ter), NCI-TCGA Cosmic COSV5073, cosmic curated COSV50736, CADD 33.00, Variant assessed as somatic; high impact.
- Y217F (p.Tyr217Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- Q220R (p.Gln220Arg), rs2541340546, ClinGen CA384363654, ClinVar RCV002597057, REVEL 0.15, MetaLR 0.28, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- S225F (p.Ser225Phe), rs1463702794, NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, gnomAD rs1463702794, REVEL 0.32, MetaLR 0.61, Variant assessed as somatic; moderate impact.
- S227R (p.Ser227Arg), rs762263587, ClinGen CA384363430, NCI-TCGA Cosmic COSV9929, ClinVar RCV004153471, AlphaMissense 0.28, MetaLR 0.32, Uncertain significance, Cardiovascular phenotype
- T229I (p.Thr229Ile), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, Ensembl rs1956952096, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- T229S (p.Thr229Ser), rs1956952096, NCI-TCGA Cosmic COSV5073, cosmic curated COSV50735, ClinGen CA384363369, REVEL 0.20, MetaLR 0.35, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- V230I (p.Val230Ile), rs543281875, ClinGen CA038350, NCI-TCGA Cosmic COSV5072, cosmic curated COSV50726, REVEL 0.24, MetaLR 0.44, Conflicting interpretations, Cardiovascular phenotype; Arrhythmogenic right ventricular cardiomyopathy; Cardi
- D232G (p.Asp232Gly), rs2541340287, ClinGen CA384363274, ClinVar RCV004125037, Uncertain significance, Cardiovascular phenotype
- D232N (p.Asp232Asn), NCI-TCGA Cosmic COSV5075, cosmic curated COSV50752, REVEL 0.25, MetaLR 0.64, Variant assessed as somatic; moderate impact.
- I234M (p.Ile234Met), rs2541340252, ClinGen CA384363193, ClinVar RCV004013218, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- P235S (p.Pro235Ser), rs2541340244, ClinGen CA384363182, ClinVar RCV004014413, ClinVar RCV005103245, REVEL 0.26, MetaLR 0.46, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9; Arrhythmogenic right ventricular c
- P238A (p.Pro238Ala), rs2541340197, ClinGen CA384363121, ClinVar RCV004012151, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- L241I (p.Leu241Ile), rs2541340118, ClinGen CA384363007, ClinVar RCV004015520, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- L241R (p.Leu241Arg), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, Variant assessed as somatic; moderate impact.
- T242A (p.Thr242Ala), rs2541340112, ClinGen CA384362980, ClinVar RCV003508551, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- Y243H (p.Tyr243His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P244H (p.Pro244His), NCI-TCGA Cosmic COSV5075, REVEL 0.23, MetaLR 0.44, Variant assessed as somatic; moderate impact.
- P244R (p.Pro244Arg), rs2541340065, ClinGen CA384362900, ClinVar RCV004519050, Uncertain significance, Cardiovascular phenotype
- G247E (p.Gly247Glu), rs767647926, ExAC rs767647926, gnomAD rs767647926, REVEL 0.28, MetaLR 0.61, Uncertain significance, Cardiovascular phenotype
- T248I (p.Thr248Ile), rs1956951485, ClinGen CA384362822, ClinVar RCV003382249, AlphaMissense 0.12, MetaLR 0.37, Uncertain significance, Cardiovascular phenotype
- S249T (p.Ser249Thr), rs1085307949, ClinGen CA384362810, ClinVar RCV003532784, AlphaMissense 0.74, MetaLR 0.74, Uncertain significance, Cardiomyopathy
- R250G (p.Arg250Gly), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99298, REVEL 0.23, MetaLR 0.51, Variant assessed as somatic; moderate impact.
- R250L (p.Arg250Leu), rs369332786, ClinGen CA038633, ClinVar RCV000694870, ClinVar RCV002388260, REVEL 0.23, MetaLR 0.45, Uncertain significance, Cardiovascular phenotype; Cardiomyopathy; Arrhythmogenic right ventricular cardi
- S251C (p.Ser251Cys), NCI-TCGA Cosmic COSV5074, cosmic curated COSV50744, Variant assessed as somatic; moderate impact.
- S251N (p.Ser251Asn), rs2541339874, ClinGen CA384362763, ClinVar RCV002717068, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- S251T (p.Ser251Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L255P (p.Leu255Pro), rs1956951118, ClinGen CA384362658, ClinVar RCV003507129, AlphaMissense 0.65, MetaLR 0.74, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- L256M (p.Leu256Met), rs1175956469, ClinGen CA384362655, ClinVar RCV003508024, AlphaMissense 0.17, MetaLR 0.59, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- E257K (p.Glu257Lys), NCI-TCGA TCGA novel, REVEL 0.44, MetaLR 0.66, Variant assessed as somatic; moderate impact.
- K258M (p.Lys258Met), NCI-TCGA TCGA novel, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- N260S (p.Asn260Ser), rs2541339766, ClinGen CA384362546, ClinVar RCV003089598, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- Y261F (p.Tyr261Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L262P (p.Leu262Pro), rs2541339735, ClinGen CA384362507, ClinVar RCV002300261, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- T263M (p.Thr263Met), rs543758984, ClinGen CA038749, NCI-TCGA Cosmic COSV5073, cosmic curated COSV50735, REVEL 0.26, MetaLR 0.42, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy; Cardiomyopathy; not provided
- A264T (p.Ala264Thr), NCI-TCGA Cosmic COSV5074, cosmic curated COSV50741, REVEL 0.18, MetaLR 0.22, Variant assessed as somatic; moderate impact.
- Q270L (p.Gln270Leu), rs2541339582, ClinGen CA384362375, ClinVar RCV004266751, Uncertain significance, Cardiovascular phenotype
- Q270R (p.Gln270Arg), rs2541339582, ClinGen CA384362376, ClinVar RCV003053607, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- R272M (p.Arg272Met), NCI-TCGA Cosmic COSV5073, cosmic curated COSV50730, Variant assessed as somatic; moderate impact.
- P273S (p.Pro273Ser), rs765756156, NCI-TCGA Cosmic COSV5073, cosmic curated COSV50734, ExAC rs765756156, REVEL 0.17, MetaLR 0.28, Variant assessed as somatic; moderate impact.
- V275M (p.Val275Met), rs2541339476, ClinGen CA384362284, ClinVar RCV003171722, REVEL 0.22, MetaLR 0.38, Uncertain significance, Cardiovascular phenotype
- P276S (p.Pro276Ser), rs201944276, ClinGen CA012521, ClinVar RCV000154802, ClinVar RCV000172583, REVEL 0.17, MetaLR 0.25, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- L277M (p.Leu277Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L277R (p.Leu277Arg), rs772827289, ClinGen CA384362239, ClinVar RCV003507193, AlphaMissense 0.08, MetaLR 0.37, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- Q278H (p.Gln278His), rs1956949832, ClinGen CA384362218, ClinVar RCV003061053, REVEL 0.18, MetaLR 0.33, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- R284K (p.Arg284Lys), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, Variant assessed as somatic; moderate impact.
- R287M (p.Arg287Met), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, Variant assessed as somatic; moderate impact.
- W290* (p.Trp290Ter), rs2541339186, ClinGen CA384362132, ClinVar RCV003508859, Pathogenic
- Q292R (p.Gln292Arg), rs1292498500, ClinGen CA384362118, ClinVar RCV003047342, NCI-TCGA TCGA novel, AlphaMissense 0.17, MetaLR 0.63, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- S294T (p.Ser294Thr), rs2541339152, ClinGen CA384362106, ClinVar RCV004016983, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- S297N (p.Ser297Asn), rs2541339091, ClinGen CA384362082, ClinVar RCV004012026, Uncertain significance, Arrhythmogenic right ventricular cardiomyopathy
- T300M (p.Thr300Met), rs553098424, ClinGen CA384362066, NCI-TCGA Cosmic COSV5074, ClinVar RCV001950468, REVEL 0.26, MetaLR 0.50, Uncertain significance, Cardiovascular phenotype; Arrhythmogenic right ventricular dysplasia 9
- R302K (p.Arg302Lys), rs2541338980, ClinGen CA384362058, ClinVar RCV003508661, Uncertain significance, Arrhythmogenic right ventricular dysplasia 9
- E303K (p.Glu303Lys), NCI-TCGA Cosmic COSV5073, cosmic curated COSV50731, Variant assessed as somatic; moderate impact.
- A304V (p.Ala304Val), NCI-TCGA Cosmic COSV9929, cosmic curated COSV99297, MetaLR 0.33, MetaSVM -0.73, Variant assessed as somatic; moderate impact.
- P306T (p.Pro306Thr), rs2541338905, ClinGen CA2825002080, ClinVar RCV004519052, REVEL 0.27, MetaLR 0.31, Likely benign, Cardiovascular phenotype
- V308C (p.Val308Cys), rs1225845438, ClinGen CA604480636, ClinVar RCV002908047, Pathogenic
Public PKP2 analysis runs
- PKP2 analysis run — PKP2 (762 variants) — completed 2026-08-10