OPTN (Optineurin) variants and mutations
OPTN (also known as Optineurin) is a human protein-coding gene encoding an optineurin protein. It serves as an adaptor in selective autophagy, vesicle trafficking, and inflammatory signaling and helps target damaged mitochondria or protein aggregates for clearance. Pathogenic variants can cause amyotrophic lateral sclerosis or certain glaucomas depending on the mechanism. This analysis covers 935 OPTN variants and mutations. Of these, 73% have computational variant effect predictions. Disease context includes open-angle glaucoma, amyotrophic lateral sclerosis, and familial amyotrophic lateral sclerosis. Example OPTN variants include M1K, S2F, and S2T.
Variant analysis overview
- Gene: OPTN
- Protein: Optineurin
- UniProt accession: Q96CV9
- Organism: Homo sapiens
- Variants analyzed: 935
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 740 unspecified-consequence records; 83 missense variants; 81 synonymous variants; 5 in-frame deletions; 7 stop-gained variants; 16 frameshift variants; 3 splice-region variants; 1 substitution
- Prediction scores: 682 variants have prediction scores (73% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: open-angle glaucoma, amyotrophic lateral sclerosis, familial amyotrophic lateral sclerosis, hereditary disease, motor neuron disorder, bone Paget disease, sarcoidosis, frontotemporal dementia, frontotemporal dementia with motor neuron disease, neurodegenerative disease, glaucoma, infection.
Protein structure and variant hotspots
- Protein features: 4 binding sites; 4 post-translational modification sites.
- PTM context: 6 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable OPTN variants
Examples include M1K, S2F, S2T, H3L, H3Y, H3R, Q4*, Q4R. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1K (p.Met1Lys), rs946553408, ClinGen CA203254115, ClinVar RCV003806665, MetaLR 0.81, MetaSVM 0.79, Uncertain significance, Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12; Glaucoma 1
- S2F (p.Ser2Phe), TOPMed rs1832936173, gnomAD rs1832936173, REVEL 0.47, CADD 26.10
- S2T (p.Ser2Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H3L (p.His3Leu), ExAC rs773681749, TOPMed rs773681749, gnomAD rs773681749, REVEL 0.28, CADD 24.00
- H3Y (p.His3Tyr), rs1554768243, ClinGen CA376026936, ClinVar RCV003781112, ClinVar RCV006276403, AlphaMissense 0.08, MetaLR 0.42, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- H3R (p.His3Arg), gnomAD 10-13109130-A-G, REVEL 0.21, CADD 21.50
- Q4* (p.Gln4Ter), cosmic curated COSV53809
- Q4R (p.Gln4Arg), gnomAD rs1441678291, REVEL 0.37, CADD 23.70
- Q4Q (p.Gln4Gln), gnomAD 10-13109134-A-G, CADD 9.94
- P5L (p.Pro5Leu), cosmic curated COSV53813
- P5R (p.Pro5Arg), rs1564354765, ClinGen CA376026953, ClinVar RCV000684859, Ensembl rs1564354765, REVEL 0.44, CADD 24.00, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- P5S (p.Pro5Ser), TOPMed rs1192626604, gnomAD rs1192626604, REVEL 0.41, CADD 21.80
- P5P (p.Pro5Pro), gnomAD 10-13109137-T-C, CADD 9.62
- L6F (p.Leu6Phe), rs747128537, ClinGen CA5410491, NCI-TCGA Cosmic COSV5381, cosmic curated COSV53810, REVEL 0.22, CADD 20.20, Uncertain significance, Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12; Glaucoma 1
- L6P (p.Leu6Pro), rs1832936570, ClinGen CA376026958, ClinVar RCV004499328, AlphaMissense 0.07, MetaLR 0.59, Uncertain significance, Inborn genetic diseases
- L6R (p.Leu6Arg), rs1832936570, ClinGen CA376026959, ClinVar RCV001108752, ClinVar RCV001108753, AlphaMissense 0.07, MetaLR 0.59, Uncertain significance, Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12
- L6V (p.Leu6Val), gnomAD 10-13109138-C-G, REVEL 0.17, CADD 16.40
- S7N (p.Ser7Asn), ESP rs370370788, ExAC rs370370788, TOPMed rs370370788, gnomAD rs370370788, REVEL 0.14, CADD 17.90
- S7R (p.Ser7Arg), gnomAD rs1244662302, REVEL 0.26, CADD 26.40
- C8G (p.Cys8Gly), gnomAD rs1437418238, REVEL 0.15, CADD 19.80
- C8Y (p.Cys8Tyr), TOPMed rs762578022, gnomAD rs762578022, REVEL 0.19, CADD 20.40
- C8S (p.Cys8Ser), gnomAD 10-13109144-T-A, REVEL 0.13, CADD 19.90
- L9F (p.Leu9Phe), Ensembl rs1832936984, REVEL 0.21, CADD 23.30
- T10S (p.Thr10Ser), Ensembl rs1044892185
- E11K (p.Glu11Lys), rs184878637, cosmic curated COSV53811, 1000Genomes rs184878637, ExAC rs184878637, REVEL 0.21, CADD 21.60, Uncertain significance, Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12; Glaucoma 1
- K12N (p.Lys12Asn), TOPMed rs1832937202
- E13V (p.Glu13Val), rs2539033411, ClinGen CA376027005, ClinVar RCV002838605, REVEL 0.25, CADD 21.00, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- E13del (p.Glu13del), rs1363880953, gnomAD 10-13109156-AAGG-, CADD 14.40
- E13* (p.Glu13Ter), gnomAD 10-13109159-G-T, CADD 36.00
- E13E (p.Glu13Glu), gnomAD 10-13109161-G-A, CADD 4.14
- D14E (p.Asp14Glu), Ensembl rs1832937262, REVEL 0.20, CADD 13.10
- D14N (p.Asp14Asn), ExAC rs759806041, TOPMed rs759806041, gnomAD rs759806041, REVEL 0.34, CADD 24.10, Uncertain significance, Inborn genetic diseases
- S15I (p.Ser15Ile), cosmic curated COSV53810
- P16A (p.Pro16Ala), rs758942502, ClinGen CA5410495, ClinVar RCV000517518, ClinVar RCV001857915, REVEL 0.47, CADD 8.59, Uncertain significance, not specified; not provided; Glaucoma 1, open angle, E
- P16L (p.Pro16Leu), gnomAD rs1346163805, REVEL 0.20, CADD 13.70
- P16T (p.Pro16Thr), ExAC rs758942502, TOPMed rs758942502, gnomAD rs758942502, Uncertain significance
- P16S (p.Pro16Ser), gnomAD 10-13109168-C-T, REVEL 0.18, CADD 9.29
- P16P (p.Pro16Pro), rs1564354813, gnomAD 10-13109170-C-T, CADD 2.61
- S17C (p.Ser17Cys), gnomAD rs1832937523, REVEL 0.27, CADD 11.40
- S17I (p.Ser17Ile), ExAC rs775446537, TOPMed rs775446537, gnomAD rs775446537, REVEL 0.29, CADD 0.01
- S17N (p.Ser17Asn), rs775446537, ClinGen CA376027031, ClinVar RCV003083441, REVEL 0.28, CADD 0.00, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- S17R (p.Ser17Arg), gnomAD 10-13109171-A-C, REVEL 0.25, CADD 8.13
- E18K (p.Glu18Lys), cosmic curated COSV53811
- E18V (p.Glu18Val), ExAC rs762818081, gnomAD rs762818081, REVEL 0.22, CADD 22.00
- S19N (p.Ser19Asn), TOPMed rs1302864896, gnomAD rs1302864896, REVEL 0.18, CADD 6.77
- T20I (p.Thr20Ile), gnomAD 10-13109181-C-T, REVEL 0.29, CADD 22.40
- T20K (p.Thr20Lys), gnomAD 10-13109181-C-A, REVEL 0.29, CADD 21.20
- G21E (p.Gly21Glu), gnomAD rs1337787932, REVEL 0.40, CADD 21.80
- G21R (p.Gly21Arg), NCI-TCGA Cosmic COSV5381, cosmic curated COSV53811, REVEL 0.36, CADD 25.30, Variant assessed as somatic; moderate impact.
- G21V (p.Gly21Val), cosmic curated COSV10941
- N22N (p.Asn22Asn), rs1832937750, gnomAD 10-13109188-T-C, CADD 8.28
- G23* (p.Gly23Ter), gnomAD rs1385369277
- G23V (p.Gly23Val), gnomAD 10-13109190-G-T, REVEL 0.63, CADD 24.20
- P24L (p.Pro24Leu), ESP rs374055453, ExAC rs374055453, TOPMed rs374055453, gnomAD rs374055453, REVEL 0.39, CADD 23.10
- P24R (p.Pro24Arg), ESP rs374055453, ExAC rs374055453, TOPMed rs374055453, gnomAD rs374055453, REVEL 0.47, CADD 22.90
- P24S (p.Pro24Ser), ExAC rs764166537, TOPMed rs764166537, gnomAD rs764166537, REVEL 0.34, CADD 19.10
- P24T (p.Pro24Thr), ExAC rs764166537, TOPMed rs764166537, gnomAD rs764166537, REVEL 0.39, CADD 18.40
- P24H (p.Pro24His), gnomAD 10-13109193-C-A, REVEL 0.32, CADD 20.70
- P24P (p.Pro24Pro), rs757085115, gnomAD 10-13109194-C-T, CADD 5.58
- P25S (p.Pro25Ser), TOPMed rs1215499993, gnomAD rs1215499993, REVEL 0.21, CADD 13.90
- P25P (p.Pro25Pro), gnomAD 10-13109197-C-A, CADD 0.91
- H26D (p.His26Asp), rs200710076, ClinGen CA5410505, cosmic curated COSV99036, ClinVar RCV002645705, REVEL 0.54, CADD 0.24, Uncertain significance, Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12; Glaucoma 1
- H26N (p.His26Asn), rs200710076, ClinGen CA5410503, ClinVar RCV002710926, ClinVar RCV004736195, REVEL 0.14, CADD 0.02, Conflicting interpretations, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- H26P (p.His26Pro), rs1832938469, ClinGen CA376027086, ClinVar RCV002409891, TOPMed rs1832938469, AlphaMissense 0.06, MetaLR 0.32, Uncertain significance, Inborn genetic diseases
- H26R (p.His26Arg), TOPMed rs1832938469, Uncertain significance, in GLC1E
- H26Y (p.His26Tyr), cosmic curated COSV10730, 1000Genomes rs200710076, ExAC rs200710076, TOPMed rs200710076, REVEL 0.20, CADD 0.12, Uncertain significance, in GLC1E
- H26T (p.His26Thr), rs753966040, gnomAD 10-13109191-AC-A, CADD 22.80
- H26H (p.His26His), rs1588433321, gnomAD 10-13109200-C-T, CADD 0.19
- L27R (p.Leu27Arg), Ensembl rs2131481036
- L27V (p.Leu27Val), gnomAD 10-13109201-C-G, REVEL 0.20, CADD 10.80
- L27L (p.Leu27Leu), gnomAD 10-13109201-C-T, CADD 5.77
- A28S (p.Ala28Ser), cosmic curated COSV53810
- H29P (p.His29Pro), Ensembl rs2131481045
- H29Q (p.His29Gln), NCI-TCGA TCGA novel, REVEL 0.16, CADD 14.70, Variant assessed as somatic; moderate impact.
- H29Y (p.His29Tyr), TOPMed rs1344210124, gnomAD rs1344210124, REVEL 0.21, CADD 19.90
- P30T (p.Pro30Thr), cosmic curated COSV10502
- P30S (p.Pro30Ser), gnomAD 10-13109210-C-T, REVEL 0.45, CADD 22.90
- N31K (p.Asn31Lys), gnomAD 10-13109211-C-CA, CADD 27.10
- L32M (p.Leu32Met), ExAC rs779662670, TOPMed rs779662670, gnomAD rs779662670, Likely benign
- L32R (p.Leu32Arg), TOPMed rs1439974533, gnomAD rs1439974533, REVEL 0.57, CADD 26.90, Uncertain significance, Amyotrophic lateral sclerosis type 12; Primary open angle glaucoma
- L32V (p.Leu32Val), rs779662670, NCI-TCGA Cosmic COSV9953, cosmic curated COSV99537, ExAC rs779662670, AlphaMissense 0.11, MetaLR 0.64, Likely benign
- L32L (p.Leu32Leu), rs779662670, gnomAD 10-13109216-C-T, AlphaMissense 0.11, MetaLR 0.64
- D33E (p.Asp33Glu), ExAC rs773608620, TOPMed rs773608620, gnomAD rs773608620
- D33H (p.Asp33His), rs2539033570, ClinGen CA376027129, ClinVar RCV003802485, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- D33V (p.Asp33Val), ExAC rs758762753, gnomAD rs758762753, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- D33D (p.Asp33Asp), rs773608620, gnomAD 10-13109221-C-T, CADD 9.14
- T34M (p.Thr34Met), rs1197658293, ClinGen CA376027139, ClinVar RCV003797842, TOPMed rs1197658293, REVEL 0.24, CADD 21.80, Uncertain significance, Amyotrophic lateral sclerosis type 12; Primary open angle glaucoma; Glaucoma 1
- T34T (p.Thr34Thr), rs2234968, gnomAD 10-13109224-G-C, CADD 0.54
- F35F (p.Phe35Phe), rs776801271, gnomAD 10-13109227-T-C, CADD 11.70
- T36A (p.Thr36Ala), TOPMed rs1832939497
- T36T (p.Thr36Thr), rs745884191, gnomAD 10-13109230-C-G, CADD 4.90
- P37L (p.Pro37Leu), rs571954285, ClinGen CA5410513, NCI-TCGA Cosmic COSV5381, cosmic curated COSV53811, REVEL 0.47, CADD 22.00, Uncertain significance, Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12; Glaucoma 1
- P37S (p.Pro37Ser), rs888024328, Ensembl rs888024328, AlphaMissense 0.32, MetaLR 0.65, Variant assessed as somatic; moderate impact.
- P37R (p.Pro37Arg), gnomAD 10-13109228-AC-A, CADD 26.80
- P37P (p.Pro37Pro), rs367658571, gnomAD 10-13109233-G-A, CADD 2.49
- E38G (p.Glu38Gly), rs1832939717, ClinGen CA376027161, ClinVar RCV002451737, Ensembl rs1832939717, AlphaMissense 0.16, MetaLR 0.61, Uncertain significance, Inborn genetic diseases
- E38E (p.Glu38Glu), rs1177703507, gnomAD 10-13109236-G-A, CADD 9.64
- E39E (p.Glu39Glu), rs762907608, gnomAD 10-13109239-G-A, CADD 9.01
- L40R (p.Leu40Arg), Ensembl rs1554768267
- L40V (p.Leu40Val), gnomAD 10-13109240-C-G, REVEL 0.27, CADD 23.00
- L40L (p.Leu40Leu), rs768586357, gnomAD 10-13109242-G-T, CADD 8.24
- L41L (p.Leu41Leu), rs11591687, gnomAD 10-13109245-G-A, CADD 8.72
- Q42H (p.Gln42His), cosmic curated COSV53810
- Q42P (p.Gln42Pro), Ensembl rs1832940129, REVEL 0.57, CADD 23.60, Uncertain significance, Glaucoma 1, open angle, E; Primary open angle glaucoma; Amyotrophic lateral scle
- Q42Q (p.Gln42Gln), gnomAD 10-13109248-G-A, CADD 6.71
- Q43* (p.Gln43Ter), rs934287314, ClinGen CA203254276, ClinVar RCV000578674, ClinVar RCV001860012, CADD 40.00, Pathogenic
- Q43del (p.Gln43del), gnomAD 10-13109244-TGCA-, CADD 17.30
- Q43Q (p.Gln43Gln), rs1832940248, gnomAD 10-13109251-G-A, CADD 8.67
- M44I (p.Met44Ile), Ensembl rs1835878869, REVEL 0.53, CADD 24.20
- M44T (p.Met44Thr), Ensembl rs1832940309, REVEL 0.62, CADD 25.80
- M44L (p.Met44Leu), gnomAD 10-13109252-A-C, REVEL 0.54, CADD 25.70
- K45Q (p.Lys45Gln), gnomAD 10-13109255-A-C, REVEL 0.34, CADD 24.20
- E46* (p.Glu46Ter), ExAC rs767309978, TOPMed rs767309978, gnomAD rs767309978
- E46D (p.Glu46Asp), gnomAD rs1832940574, REVEL 0.36, CADD 22.50
- E46K (p.Glu46Lys), ExAC rs767309978, TOPMed rs767309978, gnomAD rs767309978, REVEL 0.31, CADD 24.80
- E46V (p.Glu46Val), ExAC rs750001433, TOPMed rs750001433, gnomAD rs750001433
- L47F (p.Leu47Phe), gnomAD 10-13109261-C-T, REVEL 0.52, CADD 25.30
- L47P (p.Leu47Pro), gnomAD 10-13109262-T-C, REVEL 0.72, CADD 29.00
- L47L (p.Leu47Leu), rs1190954219, gnomAD 10-13109263-C-T, CADD 8.24
- L48M (p.Leu48Met), Ensembl rs2131481238
- L48R (p.Leu48Arg), gnomAD rs1832940696, REVEL 0.57, CADD 27.20, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- L48L (p.Leu48Leu), gnomAD 10-13109264-C-T, CADD 9.06
- T49I (p.Thr49Ile), NCI-TCGA Cosmic COSV9953, cosmic curated COSV99537, REVEL 0.21, CADD 6.09, Variant assessed as somatic; moderate impact.
- T49S (p.Thr49Ser), gnomAD 10-13109267-A-T, REVEL 0.16, CADD 15.20
- T49T (p.Thr49Thr), rs187734249, gnomAD 10-13109269-C-T, CADD 1.35
- E50D (p.Glu50Asp), NCI-TCGA Cosmic COSV5381, cosmic curated COSV53813, Variant assessed as somatic; moderate impact., in GLC1E
- E50K (p.Glu50Lys), rs28939688, ClinGen CA118628, ClinVar RCV000007513, UniProt VAR 021538, REVEL 0.66, CADD 29.90, Pathogenic, Glaucoma 1, open angle, E
- E50R (p.Glu50Arg), gnomAD 10-13109269-CG-C, CADD 33.00
- E50* (p.Glu50Ter), gnomAD 10-13109270-G-T, CADD 44.00
- N51T (p.Asn51Thr), Ensembl rs2131481260
- N51D (p.Asn51Asp), gnomAD 10-13109273-A-G, REVEL 0.57, CADD 27.60
- H52N (p.His52Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H52Y (p.His52Tyr), rs766091193, ClinGen CA5410521, ClinVar RCV003993377, ExAC rs766091193, REVEL 0.34, CADD 25.00, Uncertain significance, not provided
- H52H (p.His52His), rs1832940971, gnomAD 10-13109278-C-T, CADD 8.15
- H52Q (p.His52Gln), gnomAD 10-13109278-C-A, REVEL 0.41, CADD 23.40
- Q53* (p.Gln53Ter), Ensembl rs1832941026
- Q53del (p.Gln53del), gnomAD 10-13109278-CCAG-, CADD 20.80
- Q53H (p.Gln53His), gnomAD 10-13109281-G-T, REVEL 0.36, CADD 25.10
- L54Q (p.Leu54Gln), rs753480064, ClinGen CA376027271, ClinVar RCV002755785, ClinVar RCV004774726, REVEL 0.74, CADD 28.90, Uncertain significance, Primary open angle glaucoma; Glaucoma 1, open angle, E; Amyotrophic lateral scle
- L54R (p.Leu54Arg), ExAC rs753480064, TOPMed rs753480064, gnomAD rs753480064, REVEL 0.76, CADD 29.00, Uncertain significance
- L54V (p.Leu54Val), Ensembl rs1554768275
- L54M (p.Leu54Met), gnomAD 10-13109282-C-A, REVEL 0.52, CADD 24.60
- K55K (p.Lys55Lys), gnomAD 10-13109287-A-G, CADD 18.10
- E56V (p.Glu56Val), gnomAD rs750177059, REVEL 0.69, CADD 33.00, Uncertain significance, Inborn genetic diseases
- E56Q (p.Glu56Gln), gnomAD 10-13109288-G-C, REVEL 0.46, CADD 33.00
- A57T (p.Ala57Thr), gnomAD 10-13110276-G-A, REVEL 0.54, CADD 24.60
- A57V (p.Ala57Val), gnomAD 10-13110277-C-T, REVEL 0.58, CADD 26.20
- A57A (p.Ala57Ala), gnomAD 10-13110278-C-T, CADD 13.50
- M58T (p.Met58Thr), gnomAD rs1271759733, REVEL 0.62, CADD 25.90
- M58V (p.Met58Val), gnomAD rs1224036514, REVEL 0.41, CADD 21.80
- M58I (p.Met58Ile), gnomAD 10-13110281-G-A, REVEL 0.39, CADD 22.70
- K59M (p.Lys59Met), Ensembl rs1832967118
- K59N (p.Lys59Asn), rs1487584331, ClinGen CA376027318, ClinVar RCV001998288, ClinVar RCV002398037, REVEL 0.46, CADD 24.80, Uncertain significance, Inborn genetic diseases; Primary open angle glaucoma; Glaucoma 1, open angle, E
- K59E (p.Lys59Glu), gnomAD 10-13110282-A-G, REVEL 0.57, CADD 27.40
- N61I (p.Asn61Ile), gnomAD 10-13110289-A-T, REVEL 0.51, CADD 26.90
- N62I (p.Asn62Ile), gnomAD 10-13110292-A-T, REVEL 0.77, CADD 28.40
- Q63E (p.Gln63Glu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- Q63K (p.Gln63Lys), Ensembl rs1588434284, REVEL 0.41, CADD 24.60
- Q63P (p.Gln63Pro), Ensembl rs10047381
- A64V (p.Ala64Val), gnomAD 10-13110298-C-T, REVEL 0.31, CADD 23.10
- A64A (p.Ala64Ala), gnomAD 10-13110299-C-G, CADD 4.53
- M65T (p.Met65Thr), rs2539036228, ClinGen CA376027358, ClinVar RCV002988839, REVEL 0.67, CADD 25.70, Uncertain significance, Glaucoma 1, open angle, E; Amyotrophic lateral sclerosis type 12; Primary open a
- G67E (p.Gly67Glu), rs959069574, ClinGen CA203255155, ClinVar RCV003069701, TOPMed rs959069574, REVEL 0.24, CADD 22.50, Uncertain significance, Primary open angle glaucoma; Amyotrophic lateral sclerosis type 12; Glaucoma 1
- G67R (p.Gly67Arg), cosmic curated COSV53810
- R68K (p.Arg68Lys), cosmic curated COSV53811, gnomAD rs1186383300, REVEL 0.57, CADD 27.00
- F69C (p.Phe69Cys), NCI-TCGA Cosmic COSV5380, cosmic curated COSV53809, Variant assessed as somatic; moderate impact.
- E70Q (p.Glu70Gln), gnomAD 10-13110315-G-C, REVEL 0.56, CADD 23.60
- E70D (p.Glu70Asp), gnomAD 10-13110317-G-T, REVEL 0.50, CADD 24.00
- E71E (p.Glu71Glu), rs1832967695, gnomAD 10-13110320-G-A, CADD 11.00
- S73L (p.Ser73Leu), rs752001857, NCI-TCGA Cosmic COSV5381, cosmic curated COSV53812, ExAC rs752001857, REVEL 0.48, CADD 24.30, Variant assessed as somatic; moderate impact.
- S73S (p.Ser73Ser), rs1430621754, gnomAD 10-13110326-G-A, CADD 2.47
- A74D (p.Ala74Asp), TOPMed rs1400982119, gnomAD rs1400982119, REVEL 0.48, CADD 25.40
- A74S (p.Ala74Ser), gnomAD 10-13110327-G-T, REVEL 0.32, CADD 24.50
- W75R (p.Trp75Arg), Ensembl rs1832967921, REVEL 0.68, CADD 29.40
- T76A (p.Thr76Ala), rs757528160, ClinGen CA5410544, ClinVar RCV002301694, ExAC rs757528160, REVEL 0.23, CADD 20.50, Uncertain significance, Amyotrophic lateral sclerosis type 12; Glaucoma 1, open angle, E; Primary open a
- T76R (p.Thr76Arg), ExAC rs781755765, gnomAD rs781755765, REVEL 0.23, CADD 16.20, Uncertain significance, Inborn genetic diseases
- T76S (p.Thr76Ser), gnomAD 10-13110333-A-T, REVEL 0.22, CADD 19.50
- T76T (p.Thr76Thr), rs750952641, gnomAD 10-13110335-A-G, CADD 10.50
- E77D (p.Glu77Asp), 1000Genomes rs531691395
- E77Q (p.Glu77Gln), gnomAD 10-13110336-G-C, REVEL 0.42, CADD 26.60
Public OPTN analysis runs
- OPTN analysis run — OPTN (935 variants) — completed 2026-08-21