GAA (Lysosomal alpha-glucosidase) variants and mutations
GAA (also known as Lysosomal alpha-glucosidase) is a human protein-coding gene encoding a lysosomal alpha-glucosidase protein. It degrades lysosomal glycogen to free glucose. Biallelic loss-of-function variants cause Pompe disease, ranging from severe infantile cardiomyopathy to later-onset progressive skeletal and respiratory muscle weakness. This analysis covers 2,158 GAA variants and mutations. Of these, 75% have computational variant effect predictions. Disease context includes Glycogen storage disease due to acid maltase deficiency, glycogen storage disease II, and glycogen storage disease due to acid maltase deficiency, infantile onset. Example GAA variants include M1I, M1L, and M1T.
Variant analysis overview
- Gene: GAA
- Protein: Lysosomal alpha-glucosidase
- UniProt accession: P10253
- Organism: Homo sapiens
- Variants analyzed: 2158
- Variant scope: all variants
- Completed: 2026-08-18
Variant and mutation evidence
- Variant composition: 1,845 unspecified-consequence records; 140 missense variants; 133 synonymous variants; 20 frameshift variants; 8 stop-gained variants; 5 in-frame deletions; 1 in-frame insertions; 4 splice-region variants; 2 substitution
- Prediction scores: 1,617 variants have prediction scores (75% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Glycogen storage disease due to acid maltase deficiency, glycogen storage disease II, glycogen storage disease due to acid maltase deficiency, infantile onset, glycogen storage disease due to acid maltase deficiency, late-onset, disorder of glycogen metabolism, type 2 diabetes mellitus, Abnormality of the cardiovascular system, diabetes mellitus, Glycogen storage disease due to glycogenin deficiency, myopathy, glycogen storage disease due to glycogen branching enzyme deficiency, Elevated circulating creatine kinase concentration.
Protein structure and variant hotspots
- Protein features: 1 domains; 4 binding sites; 7 post-translational modification sites.
- Structural context: 183 variants have structural context.
- PTM context: 8 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable GAA variants
Examples include M1I, M1L, M1T, M1V, G2*, G2A, G2E, G2R. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1I (p.Met1Ile), rs1187796945, ClinGen CA401359809, ClinVar RCV001249078, MetaLR 0.53, MetaSVM -0.17, Likely pathogenic, Glycogen storage disease, type II
- M1L (p.Met1Leu), rs786204467, ClinGen CA401359799, ClinVar RCV001265217, MetaLR 0.51, MetaSVM -0.26, Likely pathogenic, Glycogen storage disease, type II
- M1T (p.Met1Thr), rs2039024047, ClinGen CA401359804, ClinVar RCV001265227, MetaLR 0.53, MetaSVM 0.01, Pathogenic, Glycogen storage disease, type II
- M1V (p.Met1Val), rs786204467, ClinGen CA273952, ClinVar RCV000169114, ClinVar RCV005632279, MetaLR 0.51, MetaSVM -0.26, Pathogenic, Glycogen storage disease, type II
- G2* (p.Gly2Ter), rs1567825175, ClinGen CA401359822, cosmic curated COSV10016, ClinVar RCV000678477, CADD 33.00, Pathogenic
- G2A (p.Gly2Ala), rs1245992455, ClinGen CA401359825, ClinVar RCV000593249, ClinVar RCV001854074, REVEL 0.28, MetaLR 0.38, Uncertain significance, not provided; Glycogen storage disease, type II
- G2E (p.Gly2Glu), gnomAD rs1245992455, REVEL 0.28, MetaLR 0.37, Uncertain significance
- G2R (p.Gly2Arg), TOPMed rs1567825175, Pathogenic
- V3A (p.Val3Ala), rs1037603957, ClinGen CA294886445, ClinVar RCV001038315, Ensembl rs1037603957, REVEL 0.24, MetaLR 0.37, Uncertain significance, Glycogen storage disease, type II
- V3L (p.Val3Leu), gnomAD 17-80104593-G-T, REVEL 0.23, MetaLR 0.41
- R4G (p.Arg4Gly), Ensembl rs2039024420
- R4K (p.Arg4Lys), rs372147077, ClinGen CA198768, ClinVar RCV000168657, ClinVar RCV000336661, REVEL 0.25, MetaLR 0.36, Uncertain significance, not provided; Glycogen storage disease, type II
- R4S (p.Arg4Ser), gnomAD rs1168255772, REVEL 0.29, MetaLR 0.47
- H5L (p.His5Leu), cosmic curated COSV10512
- H5P (p.His5Pro), Ensembl rs1598568834
- H5H (p.His5His), gnomAD 17-80104601-C-T, CADD 2.19
- P6A (p.Pro6Ala), TOPMed rs1424116613, gnomAD rs1424116613, Uncertain significance
- P6L (p.Pro6Leu), rs771409180, ClinGen CA8814756, ClinVar RCV000592568, ClinVar RCV000694708, REVEL 0.25, MetaLR 0.39, Uncertain significance, not provided; Glycogen storage disease, type II
- P6Q (p.Pro6Gln), rs771409180, ClinGen CA401359886, ClinVar RCV000805680, ExAC rs771409180, REVEL 0.35, MetaLR 0.46, Uncertain significance, Glycogen storage disease, type II
- P6S (p.Pro6Ser), rs1424116613, ClinGen CA401359883, ClinVar RCV001887422, ClinVar RCV006352565, REVEL 0.17, MetaLR 0.44, Uncertain significance, Cardiovascular phenotype; Glycogen storage disease, type II
- P6P (p.Pro6Pro), rs774703637, gnomAD 17-80104604-G-C, CADD 0.16
- P7L (p.Pro7Leu), TOPMed rs2039024892
- P7S (p.Pro7Ser), cosmic curated COSV10645
- P7T (p.Pro7Thr), TOPMed rs1457377630, Uncertain significance, Glycogen storage disease, type II
- P7P (p.Pro7Pro), rs2143823837, gnomAD 17-80104607-C-T, CADD 5.78
- C8Y (p.Cys8Tyr), ExAC rs746437229, gnomAD rs746437229, REVEL 0.24, MetaLR 0.42
- C8F (p.Cys8Phe), gnomAD 17-80104609-G-T, REVEL 0.27, MetaLR 0.43
- S9C (p.Ser9Cys), rs1598568879, ClinGen CA401359938, ClinVar RCV000996615, TOPMed rs1598568879, AlphaMissense 0.08, MetaLR 0.52, Uncertain significance, not provided; Glycogen storage disease, type II
- S9F (p.Ser9Phe), rs1598568879, ClinGen CA401359935, ClinVar RCV001313981, TOPMed rs1598568879, AlphaMissense 0.08, MetaLR 0.52, Uncertain significance, Glycogen storage disease, type II
- S9P (p.Ser9Pro), rs886042671, ClinGen CA10604542, ClinVar RCV000345427, Ensembl rs886042671, AlphaMissense 0.06, MetaLR 0.43, Uncertain significance, not provided
- S9Y (p.Ser9Tyr), gnomAD 17-80104612-C-A, REVEL 0.41, MetaLR 0.55
- H10L (p.His10Leu), rs2143823914, ClinGen CA401359950, ClinVar RCV003836446, REVEL 0.37, MetaLR 0.39, Uncertain significance, Glycogen storage disease, type II
- H10Q (p.His10Gln), TOPMed rs2039025311
- H10R (p.His10Arg), Ensembl rs2143823914, REVEL 0.22, MetaLR 0.34
- H10Y (p.His10Tyr), gnomAD rs1435052110, REVEL 0.26, MetaLR 0.33
- H10H (p.His10His), gnomAD 17-80104616-C-T, CADD 0.93
- R11G (p.Arg11Gly), rs772394815, ClinGen CA401359956, ClinVar RCV000527097, ExAC rs772394815, REVEL 0.43, MetaLR 0.38, Uncertain significance, Glycogen storage disease, type II
- R11L (p.Arg11Leu), rs138812846, ClinGen CA8814761, ClinVar RCV001367234, 1000Genomes rs138812846, REVEL 0.39, MetaLR 0.38, Uncertain significance, Glycogen storage disease, type II
- R11Q (p.Arg11Gln), rs138812846, ClinGen CA8814760, ClinVar RCV000250396, ClinVar RCV000525907, REVEL 0.25, MetaLR 0.38, Conflicting interpretations, not provided; Glycogen storage disease, type II; not specified
- R11W (p.Arg11Trp), rs772394815, ClinGen CA8814759, ClinVar RCV000537422, ExAC rs772394815, REVEL 0.23, MetaLR 0.38, Uncertain significance, Glycogen storage disease, type II
- R11R (p.Arg11Arg), gnomAD 17-80104619-G-A, CADD 0.40
- L12F (p.Leu12Phe), ExAC rs768790266, TOPMed rs768790266
- L12P (p.Leu12Pro), ExAC rs776707342, gnomAD rs776707342, REVEL 0.62, MetaLR 0.47, Uncertain significance, not provided
- L12R (p.Leu12Arg), rs775312932, gnomAD 17-80104620-CTCCT, CADD 20.20
- L12L (p.Leu12Leu), rs200548806, gnomAD 17-80104622-C-T, CADD 0.58
- A14R (p.Ala14Arg), rs2510344258, ClinGen CA913184761, ClinVar RCV003159295, Pathogenic
- A14V (p.Ala14Val), rs1221096819, ClinGen CA401360004, ClinVar RCV001984491, TOPMed rs1221096819, REVEL 0.16, MetaLR 0.39, Uncertain significance, Glycogen storage disease, type II
- A14L (p.Ala14Leu), rs760443056, gnomAD 17-80104625-GGCCG, CADD 21.50
- A14T (p.Ala14Thr), gnomAD 17-80104626-G-A, REVEL 0.19, MetaLR 0.34
- A14A (p.Ala14Ala), rs141377453, gnomAD 17-80104628-C-G, CADD 0.59
- V15I (p.Val15Ile), rs772157487, ClinGen CA8814768, ClinVar RCV000706241, ClinVar RCV005056456, REVEL 0.17, MetaLR 0.39, Uncertain significance, not provided; Glycogen storage disease, type II
- V15F (p.Val15Phe), gnomAD 17-80104629-G-T, REVEL 0.40, MetaLR 0.43
- C16S (p.Cys16Ser), ExAC rs763027933, TOPMed rs763027933, gnomAD rs763027933, REVEL 0.33, MetaLR 0.36
- C16L (p.Cys16Leu), rs768357356, gnomAD 17-80104629-G-GT, CADD 13.50
- C16* (p.Cys16Ter), gnomAD 17-80104634-C-A, CADD 27.70
- C16W (p.Cys16Trp), gnomAD 17-80104634-C-G, REVEL 0.32, MetaLR 0.57
- C16C (p.Cys16Cys), rs202168804, gnomAD 17-80104634-C-T, CADD 1.89
- A17P (p.Ala17Pro), ExAC rs751425831, TOPMed rs751425831, gnomAD rs751425831, Uncertain significance
- A17S (p.Ala17Ser), rs751425831, ClinGen CA401360048, ClinVar RCV002043328, ExAC rs751425831, REVEL 0.17, MetaLR 0.39, Uncertain significance, Glycogen storage disease, type II
- A17T (p.Ala17Thr), rs751425831, ClinGen CA8814772, ClinVar RCV000531988, ClinVar RCV003884600, REVEL 0.28, MetaLR 0.36, Uncertain significance, Glycogen storage disease, type II; not provided
- A17V (p.Ala17Val), cosmic curated COSV56411, ESP rs150797523, ExAC rs150797523, TOPMed rs150797523, REVEL 0.20, MetaLR 0.41
- L18F (p.Leu18Phe), rs1487798738, ClinGen CA401360057, ClinVar RCV002304196, TOPMed rs1487798738, AlphaMissense 0.08, MetaLR 0.42, Uncertain significance, Glycogen storage disease, type II
- L18I (p.Leu18Ile), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10016, Variant assessed as somatic; moderate impact.
- L18del (p.Leu18del), gnomAD 17-80104636-CCCT-, CADD 10.10
- L18L (p.Leu18Leu), rs886053542, gnomAD 17-80104640-C-T, CADD 0.23
- V19L (p.Val19Leu), ESP rs200343198, ExAC rs200343198, TOPMed rs200343198, gnomAD rs200343198, REVEL 0.27, MetaLR 0.34, Uncertain significance
- V19M (p.Val19Met), rs200343198, ClinGen CA8814774, ClinVar RCV000813668, ClinVar RCV002345852, REVEL 0.38, MetaLR 0.36, Uncertain significance, Cardiovascular phenotype; not provided; Glycogen storage disease, type II
- V19A (p.Val19Ala), gnomAD 17-80104642-T-C, REVEL 0.27, MetaLR 0.42
- S20C (p.Ser20Cys), rs752449306, ClinGen CA16607527, ClinVar RCV000427881, ClinVar RCV001851081, REVEL 0.26, MetaLR 0.40, Uncertain significance, Glycogen storage disease, type II; not provided
- S20F (p.Ser20Phe), ExAC rs752449306, gnomAD rs752449306, REVEL 0.25, MetaLR 0.37, Uncertain significance
- S20T (p.Ser20Thr), rs1245858495, ClinGen CA401360089, ClinVar RCV003060969, TOPMed rs1245858495, REVEL 0.25, MetaLR 0.35, Uncertain significance, Glycogen storage disease, type II
- S20S (p.Ser20Ser), rs2039027228, gnomAD 17-80104646-C-G, CADD 2.42
- L21F (p.Leu21Phe), gnomAD 17-80104649-G-T, REVEL 0.26, MetaLR 0.57
- A22T (p.Ala22Thr), gnomAD rs1192534237, REVEL 0.23, MetaLR 0.33
- A22V (p.Ala22Val), ExAC rs773089240, gnomAD rs773089240, REVEL 0.20, MetaLR 0.35
- A22E (p.Ala22Glu), gnomAD 17-80104651-C-A, REVEL 0.41, MetaLR 0.36
- A22A (p.Ala22Ala), gnomAD 17-80104652-A-C, CADD 2.98
- T23A (p.Thr23Ala), rs2289537, ClinGen CA8814777, cosmic curated COSV10739, ClinVar RCV000731715, REVEL 0.30, MetaLR 0.35, Conflicting interpretations, not provided; Glycogen storage disease, type II
- T23I (p.Thr23Ile), rs2039027538, ClinGen CA401360134, cosmic curated COSV10739, ClinVar RCV001064957, AlphaMissense 0.12, MetaLR 0.39, Uncertain significance, Glycogen storage disease, type II
- T23N (p.Thr23Asn), cosmic curated COSV10016
- T23P (p.Thr23Pro), gnomAD 17-80104653-A-C, REVEL 0.54, MetaLR 0.35
- T23T (p.Thr23Thr), rs746351336, gnomAD 17-80104655-C-A, CADD 0.04
- A24T (p.Ala24Thr), rs139716763, ClinGen CA8814780, ClinVar RCV000266365, ClinVar RCV000631058, REVEL 0.27, MetaLR 0.38, Uncertain significance, not provided; Cardiovascular phenotype; Glycogen storage disease, type II
- A24V (p.Ala24Val), Ensembl rs967596261
- A24A (p.Ala24Ala), rs747380728, gnomAD 17-80104658-T-C, CADD 3.61
- A25V (p.Ala25Val), rs768867363, ClinGen CA8814782, ClinVar RCV000593045, ClinVar RCV002530965, REVEL 0.20, MetaLR 0.34, Uncertain significance, not provided; Glycogen storage disease, type II
- A25T (p.Ala25Thr), gnomAD 17-80104659-G-A, REVEL 0.22, MetaLR 0.39
- A25S (p.Ala25Ser), gnomAD 17-80104659-G-T, REVEL 0.21, MetaLR 0.40
- A25A (p.Ala25Ala), rs1366159150, gnomAD 17-80104661-A-G, CADD 4.21
- L26F (p.Leu26Phe), rs149761650, ClinGen CA8814783, ClinVar RCV000728232, ClinVar RCV001065556, REVEL 0.24, MetaLR 0.40, Uncertain significance, not provided; Glycogen storage disease, type II
- L26R (p.Leu26Arg), rs1385098269, ClinGen CA401360183, ClinVar RCV000690873, ClinVar RCV004619384, AlphaMissense 0.30, MetaLR 0.60, Uncertain significance, Cardiovascular phenotype; Glycogen storage disease, type II
- L26H (p.Leu26His), gnomAD 17-80104658-TGCAC, CADD 24.90
- L26L (p.Leu26Leu), rs2143824668, gnomAD 17-80104664-C-T, CADD 1.76
- L27V (p.Leu27Val), 1000Genomes rs538605208, ExAC rs538605208, gnomAD rs538605208, REVEL 0.26, MetaLR 0.35, Likely benign
- L27L (p.Leu27Leu), rs538605208, gnomAD 17-80104665-C-T, CADD 1.82
- G28E (p.Gly28Glu), cosmic curated COSV10812, TOPMed rs886042598, REVEL 0.29, AlphaMissense 0.51, Uncertain significance, Glycogen storage disease, type II
- G28R (p.Gly28Arg), Ensembl rs11540428
- G28V (p.Gly28Val), rs886042598, ClinGen CA10604460, ClinVar RCV000304860, TOPMed rs886042598, AlphaMissense 0.51, MetaLR 0.43, Uncertain significance, not provided
- G28W (p.Gly28Trp), cosmic curated COSV10016
- G28G (p.Gly28Gly), rs769733901, gnomAD 17-80104670-G-A, CADD 0.59
- H29A (p.His29Ala), rs2510344492, ClinGen CA2695200345, ClinVar RCV003461621, Likely pathogenic
- H29Y (p.His29Tyr), Ensembl rs543024942, REVEL 0.24, MetaLR 0.33
- H29H (p.His29His), rs2039028572, gnomAD 17-80104673-C-T, CADD 0.41
- L31V (p.Leu31Val), TOPMed rs1295278849, Likely benign
- L32del (p.Leu32del), rs1278892703, gnomAD 17-80104676-CCTA-, CADD 9.17
- L32I (p.Leu32Ile), gnomAD 17-80104680-C-A, REVEL 0.26, MetaLR 0.65
- H33R (p.His33Arg), rs773479616, ClinGen CA8814786, ClinVar RCV001897622, ExAC rs773479616, REVEL 0.24, MetaLR 0.37, Uncertain significance, Glycogen storage disease, type II
- H33P (p.His33Pro), gnomAD 17-80104684-A-C, REVEL 0.49, MetaLR 0.38
- H33H (p.His33His), rs144736309, gnomAD 17-80104685-T-C, CADD 0.47
- D34Y (p.Asp34Tyr), ExAC rs766452755, gnomAD rs766452755, REVEL 0.46, MetaLR 0.42
- D34G (p.Asp34Gly), gnomAD 17-80104687-A-G, REVEL 0.32, MetaLR 0.43
- D34E (p.Asp34Glu), gnomAD 17-80104688-T-A, REVEL 0.16, MetaLR 0.31
- F35L (p.Phe35Leu), TOPMed rs2039029036, REVEL 0.30, MetaLR 0.27
- F35V (p.Phe35Val), NCI-TCGA Cosmic COSV5640, cosmic curated COSV56409, Variant assessed as somatic; moderate impact.
- F35F (p.Phe35Phe), gnomAD 17-80104691-C-T, CADD 0.75
- L36M (p.Leu36Met), gnomAD 17-80104692-C-A, REVEL 0.22, MetaLR 0.41
- L36L (p.Leu36Leu), gnomAD 17-80104692-C-T, CADD 0.19
- L37V (p.Leu37Val), rs369775994, ClinGen CA8814789, ClinVar RCV000702245, ClinVar RCV001556663, REVEL 0.27, MetaLR 0.34, Uncertain significance, not provided; Glycogen storage disease, type II
- V38A (p.Val38Ala), gnomAD 17-80104699-T-C, REVEL 0.16, MetaLR 0.37
- P39L (p.Pro39Leu), rs1567825457, ClinGen CA401360282, ClinVar RCV000729535, TOPMed rs1567825457, REVEL 0.19, MetaLR 0.34, Uncertain significance, not provided
- P39S (p.Pro39Ser), ExAC rs759236536, gnomAD rs759236536, REVEL 0.20, AlphaMissense 0.10, Uncertain significance
- P39T (p.Pro39Thr), rs759236536, ClinGen CA401360278, ClinVar RCV001367724, ExAC rs759236536, AlphaMissense 0.10, MetaLR 0.45, Uncertain significance, Glycogen storage disease, type II
- P39P (p.Pro39Pro), rs1449695541, gnomAD 17-80104703-C-T, CADD 4.54
- R40* (p.Arg40Ter), rs767409395, ClinGen CA8814791, ClinVar RCV000489843, ClinVar RCV000589039, CADD 35.00, Pathogenic
- R40G (p.Arg40Gly), rs767409395, ClinGen CA401360283, cosmic curated COSV56410, ClinVar RCV001043854, REVEL 0.23, MetaLR 0.39, Uncertain significance, Glycogen storage disease, type II
- R40Q (p.Arg40Gln), rs374476196, ClinGen CA8814792, ClinVar RCV000631091, ClinVar RCV002292572, REVEL 0.26, MetaLR 0.33, Conflicting interpretations, not provided; Glycogen storage disease, type II; Cardiovascular phenotype
- L42L (p.Leu42Leu), gnomAD 17-80104710-C-T, CADD 3.54
- L42V (p.Leu42Val), gnomAD 17-80104710-C-G, REVEL 0.12, MetaLR 0.40
- L42P (p.Leu42Pro), gnomAD 17-80104711-T-C, REVEL 0.21, MetaLR 0.33
- L42R (p.Leu42Arg), gnomAD 17-80104711-T-G, REVEL 0.19, MetaLR 0.32
- S43N (p.Ser43Asn), gnomAD 17-80104714-G-A, REVEL 0.21, MetaLR 0.38
- S43T (p.Ser43Thr), gnomAD 17-80104714-G-C, REVEL 0.19, MetaLR 0.38
- S43S (p.Ser43Ser), gnomAD 17-80104715-T-C, CADD 0.29
- G44D (p.Gly44Asp), ExAC rs550609502, TOPMed rs550609502, gnomAD rs550609502, REVEL 0.27, MetaLR 0.38, Uncertain significance
- G44V (p.Gly44Val), rs550609502, ClinGen CA8814793, cosmic curated COSV10609, ClinVar RCV000278138, REVEL 0.24, MetaLR 0.40, Uncertain significance, Glycogen storage disease, type II
- G44G (p.Gly44Gly), rs2143825106, gnomAD 17-80104718-C-T, CADD 1.06
- S45A (p.Ser45Ala), rs1322709296, ClinGen CA401360312, ClinVar RCV001235043, gnomAD rs1322709296, AlphaMissense 0.07, MetaLR 0.35, Uncertain significance, Glycogen storage disease, type II
- S45C (p.Ser45Cys), gnomAD rs1179395024, REVEL 0.26, MetaLR 0.42, Uncertain significance
- S45F (p.Ser45Phe), rs1179395024, ClinGen CA401360317, ClinVar RCV001359778, gnomAD rs1179395024, REVEL 0.24, MetaLR 0.41, Uncertain significance, Glycogen storage disease, type II
- S45P (p.Ser45Pro), gnomAD rs1322709296, REVEL 0.23, AlphaMissense 0.07, Uncertain significance
- S46F (p.Ser46Phe), gnomAD rs1470811257, REVEL 0.23, MetaLR 0.47
- S46P (p.Ser46Pro), rs777215354, cosmic curated COSV10883, UniProt VAR 068564, ExAC rs777215354, REVEL 0.48, MetaLR 0.37, Likely benign, Glycogen storage disease, type II
- S46S (p.Ser46Ser), rs753375900, gnomAD 17-80104724-C-T, CADD 2.26
- P47S (p.Pro47Ser), TOPMed rs969541657, gnomAD rs969541657, REVEL 0.26, MetaLR 0.33
- V48D (p.Val48Asp), gnomAD 17-80104729-T-A, REVEL 0.28, MetaLR 0.35
- V48V (p.Val48Val), rs1055575232, gnomAD 17-80104730-C-T, CADD 0.17
- L49L (p.Leu49Leu), rs915625623, gnomAD 17-80104733-G-A, CADD 1.12
- E50* (p.Glu50Ter), rs1555598609, ClinGen CA401360341, ClinVar RCV001207918, Ensembl rs1555598609, AlphaMissense 0.07, MetaLR 0.40, Pathogenic
- E50G (p.Glu50Gly), Ensembl rs2143825322
- E50K (p.Glu50Lys), rs1555598609, ClinGen CA401360339, ClinVar RCV000548222, Ensembl rs1555598609, AlphaMissense 0.07, MetaLR 0.40, Uncertain significance, Glycogen storage disease, type II
- E51G (p.Glu51Gly), TOPMed rs980788190, gnomAD rs980788190, REVEL 0.26, MetaLR 0.38
- E51K (p.Glu51Lys), rs2039030436, ClinGen CA401360347, ClinVar RCV001907344, TOPMed rs2039030436, REVEL 0.31, MetaLR 0.43, Uncertain significance, Glycogen storage disease, type II
- E51Q (p.Glu51Gln), gnomAD 17-80104737-G-C, REVEL 0.27, MetaLR 0.45
- T52A (p.Thr52Ala), Ensembl rs2143825352
- T52P (p.Thr52Pro), Ensembl rs2143825352
- H53N (p.His53Asn), ESP rs375154762, ExAC rs375154762, TOPMed rs375154762, gnomAD rs375154762, REVEL 0.17, MetaLR 0.33
- H53Q (p.His53Gln), rs2143825464, ClinGen CA401360364, ClinVar RCV002756165, REVEL 0.19, MetaLR 0.42, Uncertain significance, Glycogen storage disease, type II
- H53R (p.His53Arg), rs780554430, ClinGen CA8814797, ClinVar RCV003143452, ExAC rs780554430, REVEL 0.30, MetaLR 0.40, Uncertain significance, not provided
- H53P (p.His53Pro), rs1027029347, gnomAD 17-80104740-ACT-A, CADD 16.30
- H53H (p.His53His), rs2143825464, gnomAD 17-80104745-C-T, CADD 1.36
- P54L (p.Pro54Leu), rs768898668, ClinGen CA8814799, ClinVar RCV001248345, ExAC rs768898668, AlphaMissense 0.07, MetaLR 0.33, Uncertain significance, Glycogen storage disease, type II
- P54S (p.Pro54Ser), ExAC rs747611893
- P54T (p.Pro54Thr), ExAC rs747611893, REVEL 0.23, MetaLR 0.41
- A55V (p.Ala55Val), gnomAD 17-80104750-C-T, REVEL 0.28, MetaLR 0.45
- H56L (p.His56Leu), rs113740017, ClinGen CA294886644, ClinVar RCV001059492, Ensembl rs113740017, REVEL 0.29, MetaLR 0.37, Uncertain significance, Glycogen storage disease, type II
- H56N (p.His56Asn), rs781650771, ClinGen CA294886642, ClinVar RCV002685537, ExAC rs781650771, REVEL 0.13, MetaLR 0.39, Uncertain significance, Glycogen storage disease, type II
- H56Y (p.His56Tyr), ExAC rs781650771, TOPMed rs781650771, gnomAD rs781650771, REVEL 0.17, MetaLR 0.33, Uncertain significance
- H56D (p.His56Asp), gnomAD 17-80104752-C-G, REVEL 0.23, MetaLR 0.40
- H56H (p.His56His), rs568993202, gnomAD 17-80104754-C-T, CADD 1.51
- Q57* (p.Gln57Ter), rs1057516251, ClinGen CA16041879, ClinVar RCV000412122, ClinVar RCV003488580, Pathogenic
- Q57R (p.Gln57Arg), Ensembl rs2039031222
- Q57E (p.Gln57Glu), gnomAD 17-80104755-C-G, REVEL 0.28, MetaLR 0.37
- Q58* (p.Gln58Ter), rs201185475, ClinGen CA274104, ClinVar RCV000169263, 1000Genomes rs201185475, CADD 34.00, Pathogenic
- Q58H (p.Gln58His), TOPMed rs907769507
- Q58Q (p.Gln58Gln), gnomAD 17-80104760-G-A, CADD 3.57
- G59* (p.Gly59Ter), ExAC rs773387991, gnomAD rs773387991, CADD 34.00
- G59E (p.Gly59Glu), ExAC rs749386653, gnomAD rs749386653, REVEL 0.35, MetaLR 0.34
- G59R (p.Gly59Arg), ExAC rs773387991, gnomAD rs773387991, REVEL 0.32, MetaLR 0.42
- A60D (p.Ala60Asp), TOPMed rs1314067837, REVEL 0.30, MetaLR 0.38
- A60T (p.Ala60Thr), gnomAD rs1354152347, REVEL 0.30, MetaLR 0.36
Public GAA analysis runs
- GAA analysis run — GAA (2,158 variants) — completed 2026-08-18