CSRP3 (P50461) variants and mutations
CSRP3 (also known as P50461) is a human protein-coding gene encoding a cysteine and glycine-rich protein 3 protein. It localizes to the cardiac Z-disc and participates in mechanosensing and maintenance of sarcomere structure under mechanical load. Pathogenic variants can cause hypertrophic or dilated cardiomyopathy by disrupting cardiac structural signaling. This analysis covers 548 CSRP3 variants and mutations. Of these, 93% have computational variant effect predictions. Disease context includes dilated cardiomyopathy 1M, hypertrophic cardiomyopathy 12, and hypertrophic cardiomyopathy. Example CSRP3 variants include M1I, M1T, and P2Q.
Variant analysis overview
- Gene: CSRP3
- Protein: P50461
- UniProt accession: P50461
- Organism: Homo sapiens
- Variants analyzed: 548
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 341 unspecified-consequence records; 1 stop retained variant; 5 stop lost; 55 synonymous variants; 109 missense variants; 10 stop-gained variants; 21 frameshift variants; 3 in-frame deletions; 1 splice-region variants; 1 substitution
- Prediction scores: 511 variants have prediction scores (93% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: dilated cardiomyopathy 1M, hypertrophic cardiomyopathy 12, hypertrophic cardiomyopathy, familial isolated dilated cardiomyopathy, cardiomyopathy, Rare familial disorder with hypertrophic cardiomyopathy, Abnormality of the cardiovascular system, dilated cardiomyopathy, familial hypertrophic cardiomyopathy, hypertrophic cardiomyopathy 1, osteoarthritis, knee, osteoarthritis.
Protein structure and variant hotspots
- Protein features: 2 domains; 2 post-translational modification sites.
- Structural context: 291 variants have structural context.
- PTM context: 6 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable CSRP3 variants
Examples include M1I, M1T, P2Q, P2S, N3K, W4R, W4*, G5D. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1I (p.Met1Ile), rs2494229293, ClinGen CA379888704, ClinVar RCV003296750, Uncertain significance, Cardiovascular phenotype
- M1T (p.Met1Thr), rs2133516584, ClinGen CA379888706, ClinVar RCV001780888, MetaLR 0.45, MetaSVM -0.06, Likely pathogenic, not provided
- P2Q (p.Pro2Gln), rs762730416, ClinGen CA5916691, ClinVar RCV002943155, ExAC rs762730416, REVEL 0.46, CADD 26.00, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- P2S (p.Pro2Ser), rs2494229288, ClinGen CA379888699, ClinVar RCV002343042, REVEL 0.30, CADD 22.60, Uncertain significance, Cardiovascular phenotype
- N3K (p.Asn3Lys), Ensembl rs935934212, REVEL 0.06, CADD 17.60, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- W4R (p.Trp4Arg), rs45550635, ClinGen CA175609, ClinVar RCV000009321, ClinVar RCV000150371, REVEL 0.47, CADD 25.20, Conflicting interpretations, Sudden unexplained death; Hypertrophic cardiomyopathy; Cardiovascular phenotype
- W4* (p.Trp4Ter), gnomAD 11-19185009-C-T, REVEL 0.83, MetaLR 0.74
- G5D (p.Gly5Asp), rs2133516544, ClinGen CA379888679, ClinVar RCV001935259, Ensembl rs2133516544, AlphaMissense 0.99, MetaLR 0.60, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- G5R (p.Gly5Arg), ExAC rs769677095, TOPMed rs769677095, gnomAD rs769677095, REVEL 0.56, CADD 25.10
- G5S (p.Gly5Ser), cosmic curated COSV10723, ExAC rs769677095, TOPMed rs769677095, gnomAD rs769677095
- G6* (p.Gly6Ter), 1000Genomes rs185980145, ESP rs185980145, ExAC rs185980145, TOPMed rs185980145, CADD 37.00, Likely benign
- G6E (p.Gly6Glu), rs1431565691, ClinGen CA379888675, ClinVar RCV001065389, ClinVar RCV001170941, REVEL 0.36, CADD 24.70, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; Cardiomyopathy
- G6R (p.Gly6Arg), rs185980145, ClinGen CA175606, ClinVar RCV000150370, ClinVar RCV000623694, REVEL 0.42, CADD 25.40, Conflicting interpretations, Cardiovascular phenotype; not specified; Hypertrophic cardiomyopathy 12
- G7D (p.Gly7Asp), ExAC rs768595166, gnomAD rs768595166, MetaLR 0.54, MetaSVM 0.08
- G7V (p.Gly7Val), ExAC rs768595166, gnomAD rs768595166, REVEL 0.34, CADD 24.00
- A8E (p.Ala8Glu), cosmic curated COSV56389
- A8T (p.Ala8Thr), rs45531937, ClinGen CA5916686, cosmic curated COSV99788, ClinVar RCV000464452, REVEL 0.09, CADD 18.80, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; not provided
- K9T (p.Lys9Thr), rs1352827887, ClinGen CA379888660, ClinVar RCV000554657, ClinVar RCV003327422, REVEL 0.44, CADD 23.40, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- C10R (p.Cys10Arg), rs2133516498, ClinGen CA379888654, ClinVar RCV001989598, ClinVar RCV004045456, REVEL 0.98, CADD 26.90, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; Cardiovascular phenot
- C10Y (p.Cys10Tyr), rs141980088, ClinGen CA5916685, ClinVar RCV000698091, ClinVar RCV002440492, REVEL 0.98, CADD 25.40, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- G11E (p.Gly11Glu), rs1196538543, ClinGen CA379888644, ClinVar RCV000685705, TOPMed rs1196538543, REVEL 0.53, CADD 23.50, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- G11V (p.Gly11Val), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99788, REVEL 0.48, CADD 23.50, Variant assessed as somatic; moderate impact.
- G11G (p.Gly11Gly), gnomAD 11-19192416-T-C, CADD 8.79
- A12D (p.Ala12Asp), NCI-TCGA TCGA novel, MetaLR 0.86, MetaSVM 0.81, Variant assessed as somatic; moderate impact.
- A12G (p.Ala12Gly), rs1188954940, ClinGen CA379888638, ClinVar RCV003787598, TOPMed rs1188954940, REVEL 0.49, CADD 24.40, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- A12T (p.Ala12Thr), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99788, REVEL 0.52, CADD 23.40, Variant assessed as somatic; moderate impact.
- A12V (p.Ala12Val), gnomAD 11-19192414-G-A, REVEL 0.42, MetaLR 0.62
- C13R (p.Cys13Arg), rs1257113692, ClinGen CA379888635, ClinVar RCV001890517, ClinVar RCV002361158, REVEL 0.98, CADD 27.60, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- C13S (p.Cys13Ser), TOPMed rs1257113692, gnomAD rs1257113692, REVEL 0.98, CADD 26.30, Uncertain significance
- C13Y (p.Cys13Tyr), rs182726860, ClinGen CA5916684, ClinVar RCV003789448, ClinVar RCV005230571, REVEL 0.98, CADD 25.70, Uncertain significance, not provided; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- E14D (p.Glu14Asp), ExAC rs756368977, gnomAD rs756368977
- E14Q (p.Glu14Gln), rs777883490, ClinGen CA5916683, ClinVar RCV000653692, ClinVar RCV002325314, REVEL 0.32, CADD 16.40, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- E14E (p.Glu14Glu), rs756368977, gnomAD 11-19192407-T-C, CADD 1.70
- K15E (p.Lys15Glu), rs992234249, ClinGen CA218634859, ClinVar RCV002654713, ClinVar RCV004072034, REVEL 0.69, CADD 26.00, Uncertain significance, Cardiovascular phenotype; Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy
- K15R (p.Lys15Arg), TOPMed rs1308434550, gnomAD rs1308434550, REVEL 0.42, CADD 22.50, Uncertain significance, not specified; Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- K15K (p.Lys15Lys), rs1850631016, gnomAD 11-19192404-C-T, CADD 9.71
- T16I (p.Thr16Ile), rs397516857, ClinGen CA134906, ClinVar RCV000037785, Ensembl rs397516857, AlphaMissense 0.56, MetaLR 0.85, Uncertain significance, not specified
- T16S (p.Thr16Ser), rs1565053147, ClinGen CA379888613, ClinVar RCV000710022, Ensembl rs1565053147, AlphaMissense 0.26, MetaLR 0.65, Likely pathogenic, Primary dilated cardiomyopathy
- T16T (p.Thr16Thr), gnomAD 11-19192401-G-T, CADD 0.49
- T16N (p.Thr16Asn), gnomAD 11-19192402-G-T, REVEL 0.41, MetaLR 0.74
- V17D (p.Val17Asp), rs1060500131, ClinGen CA16613283, ClinVar RCV000471088, Ensembl rs1060500131, AlphaMissense 1.00, MetaLR 0.91, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- V17I (p.Val17Ile), rs767932680, ClinGen CA5916680, cosmic curated COSV56389, ClinVar RCV000614107, REVEL 0.49, CADD 24.90, Uncertain significance, CSRP3-related disorder; Cardiovascular phenotype; Hypertrophic cardiomyopathy 12
- V17M (p.Val17Met), rs776444956, gnomAD 11-19192393-TGGTA, CADD 32.00
- V17V (p.Val17Val), gnomAD 11-19192398-G-T, CADD 7.35
- Y18T (p.Tyr18Thr), rs759305806, gnomAD 11-19192396-TA-T, CADD 28.70
- Y18Q (p.Tyr18Gln), rs1336937886, gnomAD 11-19192398-G-GAA, CADD 28.30
- H19D (p.His19Asp), rs375525973, ClinGen CA5916678, ClinVar RCV003798554, ESP rs375525973, REVEL 0.67, CADD 24.60, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- H19H (p.His19His), rs1310682798, gnomAD 11-19192392-A-G, CADD 1.07
- A20A (p.Ala20Ala), gnomAD 11-19192389-T-C, CADD 5.36
- A20V (p.Ala20Val), gnomAD 11-19192390-G-A, REVEL 0.64, MetaLR 0.86
- E22* (p.Glu22Ter), rs1354475812, ClinGen CA379888575, ClinVar RCV002356276, NCI-TCGA Cosmic COSV5638, AlphaMissense 0.98, MetaLR 0.67, Uncertain significance
- E22K (p.Glu22Lys), gnomAD rs1354475812
- I23M (p.Ile23Met), gnomAD 11-19192380-G-C, REVEL 0.44, MetaLR 0.53
- I23I (p.Ile23Ile), gnomAD 11-19192380-G-T, CADD 11.80
- Q24H (p.Gln24His), rs1590106178, ClinGen CA379888556, ClinVar RCV003167980, Ensembl rs1590106178, AlphaMissense 0.75, MetaLR 0.86, Uncertain significance, Cardiovascular phenotype
- Q24* (p.Gln24Ter), rs1590102843, gnomAD 11-19185037-G-A, CADD 8.10, SIFT 0.41
- Q24Q (p.Gln24Gln), gnomAD 11-19192377-C-T, CADD 9.42
- Q24R (p.Gln24Arg), gnomAD 11-19192378-T-C, REVEL 0.66, MetaLR 0.83
- C25F (p.Cys25Phe), 1000Genomes rs190182843, ExAC rs190182843, TOPMed rs190182843, gnomAD rs190182843, REVEL 0.88, CADD 26.70
- C25S (p.Cys25Ser), rs2133516363, ClinGen CA379888554, ClinVar RCV001907411, Ensembl rs2133516363, REVEL 0.74, CADD 24.40, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- C25C (p.Cys25Cys), rs1328153568, gnomAD 11-19192374-G-A, CADD 12.40
- N26D (p.Asn26Asp), rs1408098337, ClinGen CA379888546, ClinVar RCV001293157, ClinVar RCV001879973, REVEL 0.35, CADD 20.50, Conflicting interpretations, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; Hypertrophic cardiomy
- N26K (p.Asn26Lys), rs909246685, ClinGen CA218634835, ClinVar RCV003795972, TOPMed rs909246685, REVEL 0.31, CADD 9.81, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- N26S (p.Asn26Ser), rs778512127, gnomAD 11-19186303-T-C, CADD 9.56, SIFT 1.00
- N26N (p.Asn26Asn), gnomAD 11-19192371-A-G, CADD 5.19
- G27A (p.Gly27Ala), gnomAD rs1416096419, REVEL 0.80, CADD 23.60
- G27E (p.Gly27Glu), cosmic curated COSV56390
- R28G (p.Arg28Gly), rs2494229022, ClinGen CA379888534, ClinVar RCV003231754, REVEL 0.44, CADD 22.70, Uncertain significance, not provided
- S29G (p.Ser29Gly), ExAC rs765951170, TOPMed rs765951170, gnomAD rs765951170, REVEL 0.69, CADD 31.00
- S29N (p.Ser29Asn), rs372717179, ClinGen CA335100, ClinVar RCV000200582, ClinVar RCV001704876, REVEL 0.53, CADD 25.10, Uncertain significance, not provided; Cardiovascular phenotype; Hypertrophic cardiomyopathy 12
- S29R (p.Ser29Arg), ExAC rs765951170, TOPMed rs765951170, gnomAD rs765951170, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- F30L (p.Phe30Leu), rs2133516315, ClinGen CA379888521, ClinVar RCV001945394, ClinVar RCV003375439, REVEL 0.86, CADD 28.00, Uncertain significance, Cardiovascular phenotype; not provided; Hypertrophic cardiomyopathy 12
- F30S (p.Phe30Ser), rs1184610308, ClinGen CA379888518, ClinVar RCV002224491, gnomAD rs1184610308, REVEL 0.87, CADD 30.00, Uncertain significance, not provided
- F30F (p.Phe30Phe), rs772727223, gnomAD 11-19192359-G-A, CADD 12.40
- H31Q (p.His31Gln), rs863225265, ClinGen CA279625, ClinVar RCV000201925, ClinVar RCV001231161, REVEL 0.90, CADD 24.60, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- H31R (p.His31Arg), TOPMed rs1850629397, MetaLR 0.97, MetaSVM 1.09
- H31Y (p.His31Tyr), gnomAD 11-19192358-G-A, REVEL 0.95, MetaLR 0.97
- K32N (p.Lys32Asn), cosmic curated COSV56389
- K32R (p.Lys32Arg), rs2133516292, ClinGen CA379888503, ClinVar RCV001552173, ClinVar RCV005209547, AlphaMissense 0.11, MetaLR 0.62, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12; not provided
- K32K (p.Lys32Lys), rs1565053085, gnomAD 11-19192353-C-T, CADD 13.80
- T33M (p.Thr33Met), rs758947977, ClinGen CA5916672, NCI-TCGA Cosmic COSV9978, cosmic curated COSV99788, REVEL 0.36, CADD 22.50, Uncertain significance, not provided; Cardiovascular phenotype; Dilated cardiomyopathy 1M
- T33T (p.Thr33Thr), rs147549410, gnomAD 11-19192350-C-A, CADD 9.18
- C34R (p.Cys34Arg), TOPMed rs1468073066, REVEL 0.96, CADD 29.40
- C34C (p.Cys34Cys), rs1453763960, gnomAD 11-19192347-A-G, CADD 9.20
- C34Y (p.Cys34Tyr), gnomAD 11-19192348-C-T, REVEL 0.94, MetaLR 0.96
- F35F (p.Phe35Phe), gnomAD 11-19192344-G-A, CADD 11.30
- H36Y (p.His36Tyr), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99788, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- H36Q (p.His36Gln), gnomAD 11-19192341-G-T, REVEL 0.35, MetaLR 0.50
- H36L (p.His36Leu), gnomAD 11-19192342-T-A, REVEL 0.24, MetaLR 0.31
- C37* (p.Cys37Ter), rs1850628800, ClinGen CA379888465, cosmic curated COSV56390, ClinVar RCV001170940, CADD 42.00, Pathogenic
- C37F (p.Cys37Phe), gnomAD rs1850628850, REVEL 0.96, CADD 32.00
- C37G (p.Cys37Gly), rs776468900, ClinGen CA379888469, ClinVar RCV000694326, ExAC rs776468900, AlphaMissense 0.99, MetaLR 0.99, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- C37R (p.Cys37Arg), rs776468900, ClinGen CA5916670, ClinVar RCV001973894, ClinVar RCV004591677, REVEL 0.94, AlphaMissense 0.99, Uncertain significance, not provided; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- C37S (p.Cys37Ser), rs760600548, gnomAD 11-19192338-GC-G, CADD 32.00
- M38I (p.Met38Ile), ExAC rs769986102, TOPMed rs769986102, gnomAD rs769986102, REVEL 0.48, CADD 23.10, Uncertain significance, Cardiovascular phenotype
- M38L (p.Met38Leu), ExAC rs768436996, gnomAD rs768436996
- M38T (p.Met38Thr), rs796360127, ClinGen CA218633685, ClinVar RCV000653695, gnomAD rs796360127, REVEL 0.48, CADD 22.30, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- A39D (p.Ala39Asp), rs748417030, ClinGen CA335103, ClinVar RCV000183334, ClinVar RCV001852350, REVEL 0.52, CADD 22.30, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- A39G (p.Ala39Gly), rs748417030, ClinGen CA5916644, ClinVar RCV001243536, ExAC rs748417030, REVEL 0.34, CADD 22.40, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; Cardiovascular phenot
- A39V (p.Ala39Val), ExAC rs748417030, TOPMed rs748417030, gnomAD rs748417030, REVEL 0.35, CADD 18.20, Uncertain significance
- A39A (p.Ala39Ala), gnomAD 11-19188300-G-A, CADD 10.40
- C40G (p.Cys40Gly), rs920763927, ClinGen CA218633676, ClinVar RCV003324470, Ensembl rs920763927, AlphaMissense 0.99, MetaLR 0.98, Uncertain significance, not specified
- C40Y (p.Cys40Tyr), rs1590104486, ClinGen CA379888440, ClinVar RCV000821461, Ensembl rs1590104486, AlphaMissense 1.00, MetaLR 0.99, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- C40C (p.Cys40Cys), rs112884796, gnomAD 11-19188297-G-A, CADD 10.60
- C40F (p.Cys40Phe), gnomAD 11-19188298-C-A, REVEL 0.98, MetaLR 0.99
- R41K (p.Arg41Lys), Ensembl rs1850562255, REVEL 0.45, CADD 19.50
- R41Q (p.Arg41Gln), rs142832902, gnomAD 11-19186336-C-T, CADD 0.59, SIFT 0.56
- R41S (p.Arg41Ser), gnomAD 11-19188294-C-G, REVEL 0.69, MetaLR 0.65
- R41R (p.Arg41Arg), rs1590104476, gnomAD 11-19188294-C-T, CADD 9.16, SIFT 0.12
- K42fsX, rs886041190, Pathogenic
- A43S (p.Ala43Ser), rs1174058654, ClinGen CA379888418, ClinVar RCV001036949, TOPMed rs1174058654, AlphaMissense 0.24, MetaLR 0.40, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- A43T (p.Ala43Thr), cosmic curated COSV56388, TOPMed rs1174058654, gnomAD rs1174058654, REVEL 0.50, AlphaMissense 0.24, Uncertain significance
- A43G (p.Ala43Gly), rs146290726, gnomAD 11-19186330-G-C, CADD 7.58, SIFT 0.47
- A43V (p.Ala43Val), rs146290726, gnomAD 11-19186330-G-A, CADD 7.79, SIFT 1.00
- L44P (p.Leu44Pro), rs104894205, ClinGen CA119913, ClinVar RCV000009323, ClinVar RCV000037770, REVEL 0.98, CADD 28.00, Conflicting interpretations, Cardiovascular phenotype; not specified; Dilated cardiomyopathy 1M
- L44V (p.Leu44Val), gnomAD rs1485902768, REVEL 0.91, CADD 25.00
- L44S (p.Leu44Ser), rs779874019, gnomAD 11-19186324-A-G, CADD 6.45, SIFT 0.85
- L44* (p.Leu44Ter), gnomAD 11-19186324-A-T, CADD 5.99, SIFT 0.15
- D45E (p.Asp45Glu), cosmic curated COSV56390, gnomAD rs1213174274, REVEL 0.74, CADD 22.50
- D45N (p.Asp45Asn), rs894467251, ClinGen CA218633669, cosmic curated COSV10956, ClinVar RCV003054638, AlphaMissense 0.96, MetaLR 0.81, Uncertain significance, Cardiovascular phenotype; Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy
- D45D (p.Asp45Asp), rs1213174274, gnomAD 11-19188282-G-A, CADD 7.89, SIFT 0.00
- S46C (p.Ser46Cys), rs137852765, ClinGen CA379888401, ClinVar RCV002383663, AlphaMissense 1.00, MetaLR 0.87, Uncertain significance, Cardiovascular phenotype
- S46G (p.Ser46Gly), rs137852765, ClinGen CA379888402, ClinVar RCV003791227, REVEL 0.81, AlphaMissense 1.00, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- S46N (p.Ser46Asn), cosmic curated COSV10801, MetaLR 0.85, MetaSVM 0.84, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- S46R (p.Ser46Arg), cosmic curated COSV56389, ExAC rs747363563, TOPMed rs747363563, gnomAD rs747363563, REVEL 0.93, AlphaMissense 1.00, Conflicting interpretations, Cardiovascular phenotype; not specified; Dilated cardiomyopathy 1M
- S46I (p.Ser46Ile), gnomAD 11-19188280-C-A, REVEL 0.83, MetaLR 0.86
- T47A (p.Thr47Ala), Ensembl rs1590104451
- T47M (p.Thr47Met), rs397516851, ClinGen CA134866, NCI-TCGA Cosmic COSV9978, cosmic curated COSV99788, REVEL 0.76, CADD 26.00, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- T47T (p.Thr47Thr), rs758842207, gnomAD 11-19188276-C-T, CADD 4.66, SIFT 0.01
- T47R (p.Thr47Arg), gnomAD 11-19188277-G-C, REVEL 0.83, MetaLR 0.85
- T48I (p.Thr48Ile), rs1850561050, ClinGen CA379888386, ClinVar RCV001342366, Ensembl rs1850561050, REVEL 0.82, AlphaMissense 0.91, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- T48K (p.Thr48Lys), rs1850561050, ClinGen CA379888388, ClinVar RCV001976617, Ensembl rs1850561050, AlphaMissense 0.91, MetaLR 0.90, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- T48A (p.Thr48Ala), gnomAD 11-19188275-T-C, REVEL 0.83, MetaLR 0.83
- V49I (p.Val49Ile), gnomAD rs1850561000, REVEL 0.41, CADD 18.90
- V49V (p.Val49Val), rs576346189, gnomAD 11-19188270-G-T, CADD 0.05
- A50E (p.Ala50Glu), rs139805841, ClinGen CA218633654, ClinVar RCV001203484, ClinVar RCV001550926, REVEL 0.81, CADD 24.50, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; not provided
- A50T (p.Ala50Thr), rs145300736, ClinGen CA134872, cosmic curated COSV56390, ClinVar RCV000037773, REVEL 0.57, CADD 17.90, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; not specified
- A50V (p.Ala50Val), rs139805841, ClinGen CA5916639, ClinVar RCV001233724, ClinVar RCV002393586, REVEL 0.67, CADD 24.60, Uncertain significance, not provided; Cardiovascular phenotype; Hypertrophic cardiomyopathy 12
- A50A (p.Ala50Ala), rs7124801, gnomAD 11-19188267-C-T, CADD 0.07, SIFT 0.00
- A51D (p.Ala51Asp), rs397516853, ClinGen CA134878, ClinVar RCV000037775, ClinVar RCV000788118, REVEL 0.49, CADD 17.30, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- A51G (p.Ala51Gly), ExAC rs397516853, TOPMed rs397516853, gnomAD rs397516853, REVEL 0.44, CADD 19.80, Uncertain significance
- A51S (p.Ala51Ser), rs1850560688, ClinGen CA379888374, ClinVar RCV001302724, Ensembl rs1850560688, AlphaMissense 0.23, MetaLR 0.46, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- A51V (p.Ala51Val), ExAC rs397516853, TOPMed rs397516853, gnomAD rs397516853, REVEL 0.43, CADD 18.20, Uncertain significance
- H52L (p.His52Leu), ExAC rs767326021, TOPMed rs767326021, gnomAD rs767326021, REVEL 0.74, AlphaMissense 0.81
- H52P (p.His52Pro), rs767326021, ClinGen CA379888370, ClinVar RCV002947483, AlphaMissense 0.81, MetaLR 0.64, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- H52Q (p.His52Gln), rs1020735963, Ensembl rs1020735963, ClinGen CA379888368, ClinVar RCV002273641, AlphaMissense 0.98, MetaLR 0.81, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; not provided
- H52R (p.His52Arg), ExAC rs767326021, TOPMed rs767326021, gnomAD rs767326021
- H52Y (p.His52Tyr), rs1590104432, ClinGen CA379888373, ClinVar RCV000788729, ClinVar RCV001856228, AlphaMissense 0.94, MetaLR 0.85, Uncertain significance, not provided; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- H52H (p.His52His), gnomAD 11-19188261-A-G, CADD 0.56, SIFT 0.00
- E53D (p.Glu53Asp), rs1253887422, ClinGen CA379888361, ClinVar RCV001982529, ClinVar RCV005542606, REVEL 0.29, CADD 7.70, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- E53K (p.Glu53Lys), rs2494223594, ClinGen CA379888367, ClinVar RCV003810472, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- E53Q (p.Glu53Gln), cosmic curated COSV10723
- S54L (p.Ser54Leu), rs759455306, ClinGen CA5916634, ClinVar RCV002401040, ClinVar RCV005227731, REVEL 0.74, CADD 22.10, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; Cardiovascular phenot
- S54N (p.Ser54Asn), rs1394465819, gnomAD 11-19186291-C-T, CADD 9.48, SIFT 0.66
- S54* (p.Ser54Ter), gnomAD 11-19188252-CTCCG, CADD 28.50
- S54S (p.Ser54Ser), rs112848043, gnomAD 11-19188255-C-T, CADD 0.16, SIFT 0.04
- E55G (p.Glu55Gly), rs267606753, ClinGen CA218633635, ClinVar RCV001754944, Ensembl rs267606753, AlphaMissense 0.87, MetaLR 0.90, Uncertain significance, not provided
- E55K (p.Glu55Lys), rs2494223567, cosmic curated COSV56390, ClinGen CA379888354, ClinVar RCV002403529, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M; Cardiovascular phenot
- I56M (p.Ile56Met), rs767360228, ClinGen CA5916632, ClinVar RCV001215019, ClinVar RCV003373043, REVEL 0.68, CADD 22.40, Uncertain significance, Cardiovascular phenotype; Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy
- I56V (p.Ile56Val), ExAC rs770041119, gnomAD rs770041119, MetaLR 0.89, MetaSVM 0.89
- p.Ile56 Tyr57del, gnomAD 11-19188245-AGTAG, CADD 16.00
- Y57H (p.Tyr57His), ESP rs374764059, ExAC rs374764059, TOPMed rs374764059, gnomAD rs374764059, REVEL 0.81, CADD 24.30, Uncertain significance, Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy 12
- C58G (p.Cys58Gly), rs104894204, ClinGen CA119911, ClinVar RCV000009322, ClinVar RCV002399315, REVEL 0.96, CADD 25.00, Pathogenic, Cardiovascular phenotype; Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy
- C58C (p.Cys58Cys), rs1057520959, gnomAD 11-19188243-G-A, CADD 4.36, SIFT 0.00
- C58F (p.Cys58Phe), gnomAD 11-19188244-C-A, REVEL 0.95, MetaLR 0.99
- C58R (p.Cys58Arg), gnomAD 11-19188245-A-G, REVEL 0.96, MetaLR 0.99
- K59E (p.Lys59Glu), rs769003538, ClinGen CA5916630, ClinVar RCV000525402, ClinVar RCV002402417, REVEL 0.87, CADD 24.60, Uncertain significance, Cardiovascular phenotype; Dilated cardiomyopathy 1M; Hypertrophic cardiomyopathy
- K59K (p.Lys59Lys), rs1850559726, gnomAD 11-19188240-C-T, CADD 2.88, SIFT 1.00
- K59N (p.Lys59Asn), gnomAD 11-19188240-C-A, REVEL 0.69, MetaLR 0.84
- V60E (p.Val60Glu), rs775072134, gnomAD 11-19186222-A-T, CADD 4.94, SIFT 0.83
- V60V (p.Val60Val), rs1486426254, gnomAD 11-19188237-C-T, CADD 4.53, SIFT 0.02
- V60G (p.Val60Gly), gnomAD 11-19188238-A-C, REVEL 0.33, MetaLR 0.57
- V60A (p.Val60Ala), gnomAD 11-19188238-A-G, REVEL 0.22, MetaLR 0.49
- V60L (p.Val60Leu), gnomAD 11-19188239-C-A, REVEL 0.27, MetaLR 0.53
- C61G (p.Cys61Gly), Ensembl rs866941870, Uncertain significance
- C61R (p.Cys61Arg), rs866941870, ClinGen CA379888314, cosmic curated COSV56389, ClinVar RCV000707101, AlphaMissense 1.00, MetaLR 0.93, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- C61Y (p.Cys61Tyr), rs2494223507, ClinGen CA379888313, ClinVar RCV003807400, Uncertain significance, Hypertrophic cardiomyopathy 12; Dilated cardiomyopathy 1M
- Y62* (p.Tyr62Ter), rs2494223496, ClinGen CA379888301, ClinVar RCV003795538, CADD 32.00, Pathogenic
- Y62C (p.Tyr62Cys), rs1850559519, ClinGen CA379888304, ClinVar RCV001808867, TOPMed rs1850559519, AlphaMissense 0.96, MetaLR 0.91, Uncertain significance, Hypertrophic cardiomyopathy 12
- G63E (p.Gly63Glu), gnomAD rs1488696683, REVEL 0.75, CADD 24.10
Public CSRP3 analysis runs
- CSRP3 analysis run — CSRP3 (548 variants) — completed 2026-08-19