CDKN1C (P49918) variants and mutations
CDKN1C (also known as P49918) is a human protein-coding gene encoding a cyclin-dependent kinase inhibitor 1C protein. It restrains embryonic and placental cell proliferation and is subject to parent-of-origin-specific genomic imprinting. Loss of maternal expression contributes to Beckwith-Wiedemann syndrome, whereas gain-of-function variants can cause growth-restriction syndromes such as IMAGe syndrome. This analysis covers 450 CDKN1C variants and mutations. Of these, 78% have computational variant effect predictions. Disease context includes Beckwith-Wiedemann syndrome, IMAGe syndrome, and neurodegenerative disease. Example CDKN1C variants include M1?, M1I, and M1T.
Variant analysis overview
- Gene: CDKN1C
- Protein: P49918
- UniProt accession: P49918
- Organism: Homo sapiens
- Variants analyzed: 450
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 200 unspecified-consequence records; 5 stop lost; 1 stop retained variant; 202 missense variants; 15 synonymous variants; 5 in-frame deletions; 17 stop-gained variants; 9 frameshift variants; 2 in-frame insertions
- Prediction scores: 353 variants have prediction scores (78% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Beckwith-Wiedemann syndrome, IMAGe syndrome, neurodegenerative disease, Alzheimer disease, multiple sclerosis, Parkinson disease, lysosomal storage disease, isolated hemihyperplasia, Beckwith-Wiedemann syndrome due to CDKN1C mutation, hereditary disease, diabetes mellitus, type 2 diabetes mellitus.
Protein structure and variant hotspots
- Protein features: 2 post-translational modification sites.
- PTM context: 11 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable CDKN1C variants
Examples include M1?, M1I, M1T, M1V, S2A, S2C, D3E, D3N. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1?, cosmic curated COSV57832
- M1I (p.Met1Ile), rs2494391518, ClinGen CA379148048, ClinVar RCV003503920, Likely pathogenic, Beckwith-Wiedemann syndrome
- M1T (p.Met1Thr), rs1848984628, ClinGen CA379148051, ClinVar RCV001302672, MetaLR 0.44, MetaSVM -0.83, Uncertain significance, Beckwith-Wiedemann syndrome
- M1V (p.Met1Val), rs1848984724, ClinGen CA379148054, ClinVar RCV001209081, MetaLR 0.44, MetaSVM -0.31, Uncertain significance, Beckwith-Wiedemann syndrome
- S2A (p.Ser2Ala), rs748680303, ClinGen CA5822254, ClinVar RCV000806732, CADD 24.50, SIFT 0.00, Uncertain significance, Beckwith-Wiedemann syndrome
- S2C (p.Ser2Cys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- D3E (p.Asp3Glu), NCI-TCGA Cosmic COSV1005, cosmic curated COSV10053, CADD 23.90, SIFT 0.01, Variant assessed as somatic; moderate impact.
- D3N (p.Asp3Asn), rs1452796504, ClinGen CA379148039, ClinVar RCV001927676, CADD 21.00, SIFT 0.54, Uncertain significance, Beckwith-Wiedemann syndrome
- A4G (p.Ala4Gly), rs201368350, ClinGen CA216367501, ClinVar RCV001340508, CADD 22.80, SIFT 0.00, Uncertain significance, Beckwith-Wiedemann syndrome
- A4T (p.Ala4Thr), rs2133786761, ClinGen CA379148033, ClinVar RCV001875681, CADD 23.60, SIFT 0.00, Uncertain significance, Beckwith-Wiedemann syndrome
- A4V (p.Ala4Val), rs201368350, ClinGen CA5822253, ClinVar RCV000628528, ClinVar RCV001814202, CADD 15.80, SIFT 1.00, Uncertain significance, Beckwith-Wiedemann syndrome; IMAGe syndrome; not provided
- L6F (p.Leu6Phe), cosmic curated COSV10053, Uncertain significance, Beckwith-Wiedemann syndrome
- L6P (p.Leu6Pro), rs201715947, ClinGen CA5822252, ClinVar RCV000456489, ClinVar RCV002523286, CADD 22.70, SIFT 0.05, Uncertain significance, Inborn genetic diseases; Beckwith-Wiedemann syndrome; IMAGe syndrome
- R7C (p.Arg7Cys), rs374634184, ClinGen CA5822251, ClinVar RCV000469288, ClinVar RCV004722759, REVEL 0.39, MetaLR 0.66, Uncertain significance, Beckwith-Wiedemann syndrome
- R7H (p.Arg7His), rs2133786706, ClinGen CA379148014, ClinVar RCV001971351, ClinVar RCV003490984, REVEL 0.34, MetaLR 0.66, Uncertain significance, not provided; Beckwith-Wiedemann syndrome
- S8R (p.Ser8Arg), cosmic curated COSV57832, CADD 22.30, SIFT 0.05
- T9I (p.Thr9Ile), rs1300493378, ClinGen CA379148002, ClinVar RCV002013909, ClinVar RCV002492347, REVEL 0.35, MetaLR 0.66, Uncertain significance, Beckwith-Wiedemann syndrome; IMAGe syndrome; Inborn genetic diseases
- T9R (p.Thr9Arg), rs1300493378, ClinGen CA379148000, ClinVar RCV003009809, AlphaMissense 0.37, MetaLR 0.30, Uncertain significance, Beckwith-Wiedemann syndrome
- S10F (p.Ser10Phe), rs1420666038, ClinGen CA379147994, ClinVar RCV001341582, CADD 23.10, SIFT 0.00, Uncertain significance, Beckwith-Wiedemann syndrome
- S10Y (p.Ser10Tyr), rs1420666038, ClinGen CA379147996, ClinVar RCV000698775, ClinVar RCV005791925, CADD 22.90, SIFT 0.00, Uncertain significance, Beckwith-Wiedemann syndrome; Inborn genetic diseases
- T11A (p.Thr11Ala), rs1564930879, ClinGen CA379147992, ClinVar RCV000703792, ClinVar RCV003483712, CADD 3.92, SIFT 1.00, Uncertain significance, Beckwith-Wiedemann syndrome
- T11M (p.Thr11Met), rs1360488872, ClinGen CA379147990, ClinVar RCV002047817, CADD 21.70, SIFT 0.01, Uncertain significance, Beckwith-Wiedemann syndrome
- M12L (p.Met12Leu), rs483352966, UniProt VAR 075200, Ensembl rs483352966, AlphaMissense 0.28, MetaLR 0.36, Uncertain significance, in BWS
- M12R (p.Met12Arg), rs2133786665, ClinGen CA379147983, ClinVar RCV002018616, AlphaMissense 0.69, MetaLR 0.47, Uncertain significance, Beckwith-Wiedemann syndrome
- M12T (p.Met12Thr), NCI-TCGA TCGA novel, Uncertain significance, in BWS
- L15P (p.Leu15Pro), rs756961090, ClinGen CA5822249, cosmic curated COSV10963, ClinVar RCV000802750, AlphaMissense 0.79, MetaLR 0.68, Uncertain significance, Beckwith-Wiedemann syndrome
- R18C (p.Arg18Cys), rs1439697461, ClinGen CA379147928, ClinVar RCV003057905, AlphaMissense 0.13, MetaLR 0.42, Uncertain significance, Beckwith-Wiedemann syndrome
- G19E (p.Gly19Glu), rs2494391115, ClinGen CA379147915, ClinVar RCV002886083, Uncertain significance, Beckwith-Wiedemann syndrome
- P22L (p.Pro22Leu), rs2494391003, ClinGen CA379147888, ClinVar RCV002796557, Uncertain significance, Beckwith-Wiedemann syndrome
- P22S (p.Pro22Ser), rs1487817041, ClinGen CA379147893, ClinVar RCV003019896, AlphaMissense 0.43, MetaLR 0.68, Uncertain significance, Beckwith-Wiedemann syndrome
- V23G (p.Val23Gly), rs2494390997, ClinGen CA379147880, ClinVar RCV002963177, Uncertain significance, Beckwith-Wiedemann syndrome
- V25M (p.Val25Met), rs758244300, ClinGen CA5822247, cosmic curated COSV10643, ClinVar RCV000794106, AlphaMissense 0.37, MetaLR 0.42, Uncertain significance, Beckwith-Wiedemann syndrome; IMAGe syndrome
- S32N (p.Ser32Asn), rs2494390738, ClinGen CA379147794, ClinVar RCV002758393, REVEL 0.15, MetaLR 0.28, Uncertain significance, Inborn genetic diseases
- L33R (p.Leu33Arg), rs2494390718, ClinGen CA379147779, ClinVar RCV003110121, Uncertain significance, not provided
- F34S (p.Phe34Ser), NCI-TCGA TCGA novel, Likely pathogenic, Beckwith-Wiedemann syndrome
- G35R (p.Gly35Arg), rs2494390648, ClinGen CA379147763, ClinVar RCV003611956, Uncertain significance, Beckwith-Wiedemann syndrome
- G35W (p.Gly35Trp), rs2494390648, ClinGen CA379147764, ClinVar RCV002807270, Uncertain significance, Beckwith-Wiedemann syndrome
- P36L (p.Pro36Leu), rs1564930749, ClinGen CA379147749, ClinVar RCV003079110, AlphaMissense 0.96, MetaLR 0.88, Uncertain significance, Inborn genetic diseases; Beckwith-Wiedemann syndrome
- P36S (p.Pro36Ser), rs2494390607, ClinGen CA379147752, ClinVar RCV003611204, Uncertain significance, Beckwith-Wiedemann syndrome
- V37L (p.Val37Leu), rs2494390561, ClinGen CA379147742, ClinVar RCV003055362, Uncertain significance, Beckwith-Wiedemann syndrome
- V37M (p.Val37Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H39N (p.His39Asn), cosmic curated COSV10963
- E40G (p.Glu40Gly), rs2494390489, ClinGen CA379147704, ClinVar RCV002782369, Uncertain significance, Inborn genetic diseases
- E40K (p.Glu40Lys), rs1564930723, ClinGen CA379147710, ClinVar RCV002604127, Ensembl rs1564930723, AlphaMissense 0.71, MetaLR 0.60, Uncertain significance, Beckwith-Wiedemann syndrome
- L42V (p.Leu42Val), rs2133786240, ClinGen CA379147684, ClinVar RCV003612467, AlphaMissense 0.77, MetaLR 0.73, Uncertain significance, Beckwith-Wiedemann syndrome
- E45* (p.Glu45Ter), rs1848977184, ClinGen CA379147654, ClinVar RCV002867481, AlphaMissense 0.66, MetaLR 0.54, Pathogenic
- Q47H (p.Gln47His), rs1060503856, ClinGen CA379147625, ClinVar RCV002838625, REVEL 0.56, MetaLR 0.68, Uncertain significance, Beckwith-Wiedemann syndrome
- Q47R (p.Gln47Arg), rs2494390317, ClinGen CA379147630, ClinVar RCV002297448, REVEL 0.36, MetaLR 0.39, Uncertain significance, Beckwith-Wiedemann syndrome
- A51T (p.Ala51Thr), rs1848975816, ClinGen CA379147598, ClinVar RCV003503455, AlphaMissense 0.99, MetaLR 0.66, Uncertain significance, Beckwith-Wiedemann syndrome
- L53P (p.Leu53Pro), rs483352968, UniProt VAR 075201, Ensembl rs483352968, AlphaMissense 1.00, MetaLR 0.60, Pathogenic, in BWS
- N54K (p.Asn54Lys), rs1230367035, ClinGen CA379147558, ClinVar RCV002304896, Uncertain significance, Beckwith-Wiedemann syndrome
- E56K (p.Glu56Lys), rs1848974871, ClinGen CA379147545, ClinVar RCV001300988, NCI-TCGA TCGA novel, AlphaMissense 0.66, MetaLR 0.54, Uncertain significance, Beckwith-Wiedemann syndrome
- D57E (p.Asp57Glu), rs777465972, ClinGen CA379147525, cosmic curated COSV57832, ClinVar RCV002051517, REVEL 0.20, MetaLR 0.29, Uncertain significance, Beckwith-Wiedemann syndrome
- R60H (p.Arg60His), cosmic curated COSV10643
- W61* (p.Trp61Ter), cosmic curated COSV57832
- Q66* (p.Gln66Ter), rs2494389957, ClinGen CA379147434, ClinVar RCV002653279, Pathogenic
- D68A (p.Asp68Ala), rs2494389922, ClinGen CA379147410, ClinVar RCV003613076, Uncertain significance, Beckwith-Wiedemann syndrome
- M69V (p.Met69Val), rs2494389907, ClinGen CA379147402, ClinVar RCV003612803, cosmic curated COSV57832, Uncertain significance, Beckwith-Wiedemann syndrome
- M69T (p.Met69Thr), gnomAD 11-2884085-A-G, CADD 4.29
- P70L (p.Pro70Leu), rs483352970, ClinGen CA216367420, ClinVar RCV001269845, ClinVar RCV003502515, AlphaMissense 1.00, MetaLR 0.99, Pathogenic/Likely pathogenic, not provided; Beckwith-Wiedemann syndrome
- R72G (p.Arg72Gly), rs2494389853, ClinGen CA379147372, ClinVar RCV002761549, Uncertain significance, Beckwith-Wiedemann syndrome
- P74S (p.Pro74Ser), rs2494389803, ClinGen CA379147348, ClinVar RCV002510088, Uncertain significance, not provided
- R76S (p.Arg76Ser), rs750526402, ClinVar RCV004590756, AlphaMissense 0.84, MetaLR 0.74, Uncertain significance, not provided
- Q78* (p.Gln78Ter), rs2133785734, ClinGen CA379147309, cosmic curated COSV57832, ClinVar RCV001382544, Pathogenic
- W79* (p.Trp79Ter), gnomAD 11-2884033-C-T, REVEL 0.66, CADD 29.90
- W79L (p.Trp79Leu), rs763529383, gnomAD 11-2884034-C-A, MetaLR 0.21, MetaSVM -0.86
- S84T (p.Ser84Thr), rs1848970951, ClinGen CA379147222, ClinVar RCV003877865, AlphaMissense 0.44, MetaLR 0.57, Uncertain significance, Beckwith-Wiedemann syndrome
- D85G (p.Asp85Gly), gnomAD 11-2884112-T-C, CADD 16.50
- S86* (p.Ser86Ter), rs897964106, ClinGen CA379147195, ClinVar RCV003030956, AlphaMissense 0.35, MetaLR 0.64, Pathogenic
- S86A (p.Ser86Ala), rs1848970693, ClinGen CA379147198, cosmic curated COSV10462, ClinVar RCV001248015, AlphaMissense 0.12, MetaLR 0.60, Uncertain significance, Beckwith-Wiedemann syndrome
- S86L (p.Ser86Leu), rs897964106, ClinGen CA379147197, ClinVar RCV003611347, gnomAD rs897964106, AlphaMissense 0.35, MetaLR 0.64, Uncertain significance, Beckwith-Wiedemann syndrome
- S86N (p.Ser86Asn), rs1314520245, gnomAD 11-2884097-C-T, CADD 9.40
- S86F (p.Ser86Phe), rs1458849556, gnomAD 11-2884130-G-A, CADD 15.10
- P88S (p.Pro88Ser), cosmic curated COSV57832
- P88L (p.Pro88Leu), rs939444064, gnomAD 11-2884124-G-A, CADD 15.80
- P88Q (p.Pro88Gln), gnomAD 11-2884124-G-T, CADD 15.10
- A89V (p.Ala89Val), rs1564928743, gnomAD 11-2884118-G-A, CADD 15.40
- A89E (p.Ala89Glu), gnomAD 11-2884118-G-T, CADD 14.30
- F90L (p.Phe90Leu), rs2133785564, ClinGen CA379147139, ClinVar RCV003033930, Uncertain significance, Beckwith-Wiedemann syndrome
- Y91C (p.Tyr91Cys), rs2494389471, ClinGen CA379147132, ClinVar RCV003329008, ClinVar RCV005310973, Uncertain significance, not provided; Inborn genetic diseases
- R92H (p.Arg92His), rs1554937506, gnomAD 11-2884106-C-T, CADD 14.20
- R92L (p.Arg92Leu), gnomAD 11-2884106-C-A, CADD 13.80
- R92K (p.Arg92Lys), rs1848882642, gnomAD 11-2884115-C-T, CADD 14.70
- R92* (p.Arg92Ter), gnomAD 11-2884116-T-A, REVEL 0.69, CADD 32.00
- T94P (p.Thr94Pro), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V95M (p.Val95Met), rs762106424, ClinGen CA5822220, NCI-TCGA Cosmic COSV5783, cosmic curated COSV57832, AlphaMissense 0.67, MetaLR 0.70, Uncertain significance, Beckwith-Wiedemann syndrome
- Q96P (p.Gln96Pro), rs1848877871, gnomAD 11-2884061-T-G, MetaLR 0.26, MetaSVM -0.87
- Q96R (p.Gln96Arg), gnomAD 11-2884061-T-C, MetaLR 0.26, MetaSVM -0.91
- Q96* (p.Gln96Ter), rs868414645, gnomAD 11-2884062-G-A, REVEL 0.28, CADD 23.80
- Q96L (p.Gln96Leu), gnomAD 11-2884109-T-A, CADD 13.10
- G98E (p.Gly98Glu), rs1398439636, ClinGen CA379147049, cosmic curated COSV10589, ClinVar RCV001897442, AlphaMissense 0.99, MetaLR 0.70, Uncertain significance, Beckwith-Wiedemann syndrome
- R99A (p.Arg99Ala), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- R99H (p.Arg99His), rs1287328131, gnomAD rs1287328131, MetaLR 0.50, MetaSVM -0.43, Uncertain significance, Beckwith-Wiedemann syndrome
- R99P (p.Arg99Pro), rs373252940, gnomAD 11-2884094-C-G, CADD 8.34
- R99L (p.Arg99Leu), gnomAD 11-2884094-C-A, CADD 7.58
- R99K (p.Arg99Lys), gnomAD 11-2884100-C-T, CADD 11.80
- R99* (p.Arg99Ter), gnomAD 11-2884101-T-A, REVEL 0.34, CADD 28.20
- C100R (p.Cys100Arg), cosmic curated COSV10053
- C100* (p.Cys100Ter), gnomAD 11-2884009-G-T, CADD 15.30
- C100F (p.Cys100Phe), rs2133779878, gnomAD 11-2884010-C-A, MetaLR 0.65, MetaSVM 0.33
- C100Y (p.Cys100Tyr), gnomAD 11-2884010-C-T, MetaLR 0.65, MetaSVM 0.33
- L102Q (p.Leu102Gln), gnomAD 11-2884103-A-T, CADD 12.90
- L102P (p.Leu102Pro), gnomAD 11-2884103-A-G, CADD 13.50
- L102R (p.Leu102Arg), gnomAD 11-2884103-A-C, CADD 13.00
- L104P (p.Leu104Pro), gnomAD 11-2884064-A-G, MetaLR 0.33, MetaSVM -0.82
- A105V (p.Ala105Val), rs2494389196, ClinGen CA379146972, ClinVar RCV002615267, Uncertain significance, Beckwith-Wiedemann syndrome
- A105G (p.Ala105Gly), gnomAD 11-2884088-G-C, CADD 6.78
- A105E (p.Ala105Glu), gnomAD 11-2884088-G-T, CADD 6.22
- P106R (p.Pro106Arg), rs1848966308, ClinVar RCV004575553, REVEL 0.21, CADD 23.80, Uncertain significance, Beckwith-Wiedemann syndrome
- P106Q (p.Pro106Gln), rs773166985, gnomAD 11-2884079-G-T, CADD 5.27
- P106L (p.Pro106Leu), rs773166985, gnomAD 11-2884079-G-A, CADD 5.83
- R107L (p.Arg107Leu), rs1235021375, gnomAD 11-2883857-AGC-A, CADD 15.60
- R107R (p.Arg107Arg), gnomAD 11-2883858-G-A, CADD 16.60
- R107H (p.Arg107His), gnomAD 11-2883859-C-T, CADD 14.50, SIFT 0.30
- R107S (p.Arg107Ser), rs552955353, gnomAD 11-2883860-G-T, CADD 17.40, SIFT 0.45
- R107C (p.Arg107Cys), rs552955353, gnomAD 11-2883860-G-A, CADD 17.70, SIFT 0.03
- R107A (p.Arg107Ala), gnomAD 11-2883863-CT-C, CADD 14.20
- R107Q (p.Arg107Gln), rs1848863397, gnomAD 11-2883874-C-T, CADD 17.70, SIFT 0.00
- R107W (p.Arg107Trp), rs1469017919, gnomAD 11-2883875-G-A, CADD 18.90, SIFT 0.00
- R107P (p.Arg107Pro), gnomAD 11-2883895-C-G, CADD 17.20, SIFT 0.13
- R107* (p.Arg107Ter), gnomAD 11-2883896-G-A, CADD 17.10
- R107K (p.Arg107Lys), rs1234859950, gnomAD 11-2884016-C-T, MetaLR 0.31, MetaSVM -0.83
- P108Q (p.Pro108Gln), gnomAD 11-2884055-G-T, MetaLR 0.39, MetaSVM -0.63
- P108L (p.Pro108Leu), rs1848877421, gnomAD 11-2884055-G-A, MetaLR 0.39, MetaSVM -0.65
- P108H (p.Pro108His), gnomAD 11-2884067-G-T, CADD 6.56
- P108R (p.Pro108Arg), rs779172459, gnomAD 11-2884067-G-C, CADD 6.68
- V109L (p.Val109Leu), rs2133785299, ClinGen CA379146932, ClinVar RCV003850145, AlphaMissense 0.14, MetaLR 0.45, Uncertain significance, Beckwith-Wiedemann syndrome
- V109A (p.Val109Ala), rs1564928644, gnomAD 11-2884070-A-G, AlphaMissense 0.09, MetaLR 0.21
- A110V (p.Ala110Val), rs2494389044, ClinGen CA379146920, ClinVar RCV003110456, Uncertain significance, Beckwith-Wiedemann syndrome
- V111A (p.Val111Ala), rs2494389018, ClinGen CA379146915, ClinVar RCV003611068, Uncertain significance, Beckwith-Wiedemann syndrome
- V111F (p.Val111Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A112T (p.Ala112Thr), NCI-TCGA TCGA novel, REVEL 0.17, CADD 14.90, Uncertain significance, Beckwith-Wiedemann syndrome
- A112V (p.Ala112Val), rs1176153874, ClinGen CA379146908, cosmic curated COSV57832, ClinVar RCV003829474, REVEL 0.16, CADD 12.00, Uncertain significance, Beckwith-Wiedemann syndrome; IMAGe syndrome
- V113W (p.Val113Trp), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- A114V (p.Ala114Val), rs2133779977, gnomAD 11-2884040-G-A, MetaLR 0.33, MetaSVM -0.78
- A114D (p.Ala114Asp), gnomAD 11-2884040-G-T, MetaLR 0.33, MetaSVM -0.69
- A114E (p.Ala114Glu), rs377216794, gnomAD 11-2884046-G-T, MetaLR 0.19, MetaSVM -0.76
- S116N (p.Ser116Asn), gnomAD 11-2884031-C-T, MetaLR 0.77, MetaSVM 0.65
- S116F (p.Ser116Phe), gnomAD 11-2884082-G-A, CADD 3.36
- S116Y (p.Ser116Tyr), rs2133780180, gnomAD 11-2884082-G-T, CADD 2.84
- P117L (p.Pro117Leu), rs1802775, gnomAD 11-2884052-G-A, MetaLR 0.34, MetaSVM -0.76
- P117H (p.Pro117His), rs1802775, gnomAD 11-2884052-G-T, MetaLR 0.41, MetaSVM -0.46
- L119V (p.Leu119Val), rs1323156745, ClinGen CA379146872, ClinVar RCV002299373, AlphaMissense 0.11, MetaLR 0.44, Uncertain significance, Beckwith-Wiedemann syndrome
- L119R (p.Leu119Arg), rs780417247, gnomAD 11-2884049-A-C, MetaLR 0.21, MetaSVM -0.90
- L119P (p.Leu119Pro), rs780417247, gnomAD 11-2884049-A-G, MetaLR 0.27, MetaSVM -0.89
- L119Q (p.Leu119Gln), gnomAD 11-2884049-A-T, MetaLR 0.21, MetaSVM -0.91
- P121S (p.Pro121Ser), rs2494388735, ClinGen CA379146857, ClinVar RCV003034279, Uncertain significance, Beckwith-Wiedemann syndrome
- P121H (p.Pro121His), rs1405293895, gnomAD 11-2884025-G-T, MetaLR 0.51, MetaSVM -0.12
- P121L (p.Pro121Leu), gnomAD 11-2884025-G-A, MetaLR 0.35, MetaSVM -0.74
- A122S (p.Ala122Ser), rs551863674, ClinGen CA379146852, ClinVar RCV002942101, AlphaMissense 0.08, MetaLR 0.41, Uncertain significance, Beckwith-Wiedemann syndrome
- A123E (p.Ala123Glu), gnomAD 11-2884019-G-T, MetaLR 0.36, MetaSVM -0.48
- A123V (p.Ala123Val), rs1848873750, gnomAD 11-2884019-G-A, MetaLR 0.36, MetaSVM -0.48
- E124K (p.Glu124Lys), cosmic curated COSV10053
- S125T (p.Ser125Thr), rs1319558011, ClinGen CA379146834, ClinVar RCV003034334, AlphaMissense 0.11, MetaLR 0.44, Uncertain significance, Beckwith-Wiedemann syndrome
- L126P (p.Leu126Pro), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G128V (p.Gly128Val), rs1848860637, gnomAD 11-2883793-C-A, CADD 18.10, SIFT 0.00
- G128C (p.Gly128Cys), rs904167456, gnomAD 11-2883794-C-A, CADD 18.80, SIFT 0.00
- G128R (p.Gly128Arg), rs904167456, gnomAD 11-2883794-C-G, CADD 19.00, SIFT 0.00
- G163del (p.Gly163del), gnomAD 11-2883812-AGCC-A, CADD 17.60
- G128G (p.Gly128Gly), gnomAD 11-2883813-G-A, CADD 18.90
- G128D (p.Gly128Asp), gnomAD 11-2883814-C-T, CADD 18.80, SIFT 0.66
- G128S (p.Gly128Ser), rs1167946710, gnomAD 11-2883815-C-T, CADD 17.30, SIFT 1.00
- G128E (p.Gly128Glu), gnomAD 11-2883844-C-T, CADD 21.40, SIFT 0.00
- G128W (p.Gly128Trp), gnomAD 11-2883845-C-A, CADD 20.40, SIFT 0.00
- G128A (p.Gly128Ala), gnomAD 11-2883880-C-G, CADD 18.10, SIFT 0.18
- L129V (p.Leu129Val), rs2494388540, ClinGen CA379146807, ClinVar RCV002801807, Uncertain significance, Beckwith-Wiedemann syndrome
- E130D (p.Glu130Asp), cosmic curated COSV10810, ExAC rs778772076, gnomAD rs778772076
- E130Q (p.Glu130Gln), rs1564930265, ClinGen CA379146801, ClinVar RCV003475634, NCI-TCGA TCGA novel, AlphaMissense 0.15, MetaLR 0.53, Uncertain significance, Beckwith-Wiedemann syndrome
- E130E (p.Glu130Glu), gnomAD 11-2884003-C-T, CADD 18.70
- E130* (p.Glu130Ter), rs1363802623, gnomAD 11-2884005-C-A, CADD 17.30
- E130K (p.Glu130Lys), rs1363802623, gnomAD 11-2884005-C-T, MetaLR 0.48, MetaSVM -0.18
- P133P (p.Pro133Pro), gnomAD 11-2883906-G-T, CADD 14.90
- P133H (p.Pro133His), gnomAD 11-2883907-G-T, CADD 16.50, SIFT 0.00
- P133R (p.Pro133Arg), rs1281208086, gnomAD 11-2883907-G-C, CADD 16.60, SIFT 0.00
- P133L (p.Pro133Leu), rs1281208086, gnomAD 11-2883907-G-A, CADD 16.80, SIFT 0.00
- P133S (p.Pro133Ser), gnomAD 11-2883908-G-A, CADD 12.70, SIFT 0.01
- P133T (p.Pro133Thr), gnomAD 11-2883908-G-T, CADD 12.50, SIFT 0.01
- P133A (p.Pro133Ala), gnomAD 11-2883908-G-C, CADD 12.60, SIFT 0.21
- P133Q (p.Pro133Gln), gnomAD 11-2884001-G-T, MetaLR 0.34, MetaSVM -0.79
- E134D (p.Glu134Asp), gnomAD 11-2883864-T-A, CADD 16.10, SIFT 0.15
Public CDKN1C analysis runs
- CDKN1C analysis run — CDKN1C (450 variants) — completed 2026-08-21