USH2A (Usherin) variants and mutations
USH2A (also known as Usherin) is a human protein-coding gene encoding an usherin protein. It helps organize extracellular and membrane structures required for cochlear hair-cell and photoreceptor function. Biallelic pathogenic variants cause Usher syndrome type 2A or nonsyndromic retinitis pigmentosa and can also produce isolated hearing loss. This analysis covers 8,895 USH2A variants and mutations. Of these, 79% have computational variant effect predictions. Disease context includes Usher syndrome type 2A, retinitis pigmentosa, and Usher syndrome. Example USH2A variants include M1V, N2D, and N2I.
Variant analysis overview
- Gene: USH2A
- Protein: Usherin
- UniProt accession: O75445
- Organism: Homo sapiens
- Variants analyzed: 8895
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 8,637 unspecified-consequence records; 102 synonymous variants; 104 missense variants; 12 in-frame deletions; 33 frameshift variants; 1 in-frame insertions; 1 stop-gained variants; 5 splice-region variants
- Prediction scores: 7,024 variants have prediction scores (79% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Usher syndrome type 2A, retinitis pigmentosa, Usher syndrome, Usher syndrome type 2, Retinal dystrophy, retinal disorder, Rare genetic deafness, hereditary disease, Cone rod dystrophy, cone-rod dystrophy, ear malformation, Abnormality of the ear.
Protein structure and variant hotspots
- Protein features: 1 transmembrane segments; 47 domains; 66 post-translational modification sites.
- Structural context: 7,304 variants have structural context.
- PTM context: 82 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable USH2A variants
Examples include M1V, N2D, N2I, N2K, N2S, C3G, C3R, C3Y. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1V (p.Met1Val), rs924627806, ClinGen CA37922164, ClinVar RCV000669526, ClinVar RCV001101305, MetaLR 0.05, MetaSVM -1.14, Likely pathogenic
- N2D (p.Asn2Asp), Ensembl rs2039693688, REVEL 0.04, CADD 1.06
- N2I (p.Asn2Ile), ExAC rs772861429, TOPMed rs772861429, gnomAD rs772861429, REVEL 0.04, CADD 6.51, Uncertain significance, not provided
- N2K (p.Asn2Lys), TOPMed rs950281688, gnomAD rs950281688, REVEL 0.06, CADD 1.82
- N2S (p.Asn2Ser), rs772861429, ClinGen CA1396871, ClinVar RCV001986860, ExAC rs772861429, REVEL 0.04, CADD 2.68, Uncertain significance, not provided
- C3G (p.Cys3Gly), TOPMed rs1007387309
- C3R (p.Cys3Arg), rs1007387309, TOPMed rs1007387309, AlphaMissense 0.08, MetaLR 0.04, Variant assessed as somatic; moderate impact.
- C3Y (p.Cys3Tyr), ExAC rs772068113, gnomAD rs772068113, REVEL 0.05, CADD 5.35, Uncertain significance, Usher syndrome type 2A
- P4L (p.Pro4Leu), TOPMed rs1345731215, gnomAD rs1345731215, REVEL 0.02, CADD 0.25
- P4Q (p.Pro4Gln), cosmic curated COSV10024, TOPMed rs1345731215, gnomAD rs1345731215, REVEL 0.02, CADD 7.51
- S7* (p.Ser7Ter), rs2527655909, ClinGen CA344905190, ClinVar RCV003579080, Pathogenic
- S7L (p.Ser7Leu), NCI-TCGA Cosmic COSV5632, cosmic curated COSV56327, MetaLR 0.01, MetaSVM -0.95, Variant assessed as somatic; moderate impact.
- L8M (p.Leu8Met), rs778803503, ClinGen CA1396869, ClinVar RCV003121415, ExAC rs778803503, REVEL 0.01, CADD 0.10, Uncertain significance, not provided
- G9D (p.Gly9Asp), Ensembl rs2102789288, REVEL 0.03, CADD 4.51
- G9R (p.Gly9Arg), cosmic curated COSV56332, ExAC rs749498075, gnomAD rs749498075, REVEL 0.03, CADD 4.06
- G9S (p.Gly9Ser), ExAC rs749498075, gnomAD rs749498075
- S10P (p.Ser10Pro), rs780210186, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10023, ExAC rs780210186, REVEL 0.03, CADD 7.77, Variant assessed as somatic; moderate impact.
- S10Y (p.Ser10Tyr), NCI-TCGA TCGA novel, MetaLR 0.02, MetaSVM -0.96, Variant assessed as somatic; moderate impact.
- F12C (p.Phe12Cys), rs2039692556, ClinGen CA344905162, ClinVar RCV003890617, Ensembl rs2039692556, REVEL 0.17, CADD 21.00, Uncertain significance, Retinal dystrophy
- F12L (p.Phe12Leu), ExAC rs756209948, TOPMed rs756209948, gnomAD rs756209948, REVEL 0.07, CADD 15.30
- F12V (p.Phe12Val), NCI-TCGA Cosmic COSV5634, cosmic curated COSV56340, MetaLR 0.03, MetaSVM -0.96, Variant assessed as somatic; moderate impact.
- L13S (p.Leu13Ser), TOPMed rs1403463697, gnomAD rs1403463697, REVEL 0.09, CADD 14.90
- F14C (p.Phe14Cys), NCI-TCGA TCGA novel, MetaLR 0.04, MetaSVM -1.02, Variant assessed as somatic; moderate impact.
- Q15* (p.Gln15Ter), rs1553258122, ClinGen CA344905143, ClinVar RCV000670151, ClinVar RCV001855538, Pathogenic
- Q15R (p.Gln15Arg), gnomAD rs1325244826, REVEL 0.01, CADD 0.03
- V16F (p.Val16Phe), ExAC rs750448122, gnomAD rs750448122, REVEL 0.07, AlphaMissense 0.09
- V16I (p.Val16Ile), rs750448122, ClinGen CA344905136, ClinVar RCV002308636, AlphaMissense 0.09, MetaLR 0.05, Uncertain significance, not specified
- I17T (p.Ile17Thr), rs942541689, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10024, gnomAD rs942541689, REVEL 0.03, CADD 0.64, Variant assessed as somatic; moderate impact.
- E18D (p.Glu18Asp), TOPMed rs1396916932, gnomAD rs1396916932, REVEL 0.09, CADD 8.75
- E18G (p.Glu18Gly), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- E18Q (p.Glu18Gln), NCI-TCGA Cosmic COSV5633, cosmic curated COSV56331, MetaLR 0.04, MetaSVM -1.03, Variant assessed as somatic; moderate impact.
- M19I (p.Met19Ile), cosmic curated COSV56366, TOPMed rs1402621522, gnomAD rs1402621522, REVEL 0.05, CADD 0.00
- M19R (p.Met19Arg), gnomAD rs1415653978, REVEL 0.07, CADD 17.10
- L20F (p.Leu20Phe), rs767611127, ClinGen CA344905104, ClinVar RCV002051240, ClinVar RCV005606976, REVEL 0.06, CADD 7.48, Uncertain significance, not provided
- I21V (p.Ile21Val), ExAC rs757708683, gnomAD rs757708683, REVEL 0.03, CADD 0.72
- F22L (p.Phe22Leu), TOPMed rs1330680909, gnomAD rs1330680909, REVEL 0.05, CADD 13.20
- A23D (p.Ala23Asp), TOPMed rs1161919436, gnomAD rs1161919436, REVEL 0.09, CADD 18.50
- A23T (p.Ala23Thr), ESP rs373342640, ExAC rs373342640, TOPMed rs373342640, gnomAD rs373342640
- A23V (p.Ala23Val), TOPMed rs1161919436, gnomAD rs1161919436, REVEL 0.05, CADD 10.10
- Y24C (p.Tyr24Cys), cosmic curated COSV56377, TOPMed rs2039691686, REVEL 0.02, CADD 2.39
- Y24H (p.Tyr24His), TOPMed rs2039691730, gnomAD rs2039691730, REVEL 0.10, CADD 15.80
- F25V (p.Phe25Val), ESP rs370619684, TOPMed rs370619684, gnomAD rs370619684, REVEL 0.02, CADD 10.60
- A26V (p.Ala26Val), cosmic curated COSV56392, ExAC rs764409229, TOPMed rs764409229, gnomAD rs764409229, REVEL 0.04, CADD 1.97
- S27L (p.Ser27Leu), Ensembl rs2039691158, MetaLR 0.04, MetaSVM -1.01
- I28M (p.Ile28Met), rs1270426964, TOPMed rs1270426964, AlphaMissense 0.09, MetaLR 0.04, Variant assessed as somatic; moderate impact.
- I28V (p.Ile28Val), rs753515909, ClinGen CA1396858, ClinVar RCV001305273, ClinVar RCV001835477, REVEL 0.02, CADD 0.00, Uncertain significance
- S29F (p.Ser29Phe), NCI-TCGA Cosmic COSV1002, NCI-TCGA Cosmic COSV5639, cosmic curated COSV56397, Variant assessed as somatic; moderate impact.
- S29T (p.Ser29Thr), rs377309313, ClinGen CA1396857, ClinVar RCV002633852, ClinVar RCV002633853, REVEL 0.01, CADD 2.65, Uncertain significance, Inborn genetic diseases; not provided; Retinitis pigmentosa 39
- S29Y (p.Ser29Tyr), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10024, NCI-TCGA Cosmic COSV5639, MetaLR 0.05, MetaSVM -1.05, Variant assessed as somatic; moderate impact.
- L30* (p.Leu30Ter), rs2527655487, ClinGen CA344905045, ClinVar RCV003464783, CADD 33.00, Pathogenic
- L30F (p.Leu30Phe), gnomAD rs763164382, REVEL 0.04, CADD 13.30
- T31A (p.Thr31Ala), rs373207201, ClinGen CA1396856, ClinVar RCV001930943, ESP rs373207201, REVEL 0.10, CADD 9.62, Uncertain significance, not provided
- T31I (p.Thr31Ile), rs750745352, ClinGen CA37922155, ClinVar RCV002854881, ClinVar RCV004691523, REVEL 0.02, CADD 14.60, Uncertain significance, Inborn genetic diseases; not provided
- T31N (p.Thr31Asn), NCI-TCGA Cosmic COSV1002, NCI-TCGA Cosmic COSV5633, cosmic curated COSV56335, MetaLR 0.03, MetaSVM -1.04, Variant assessed as somatic; moderate impact.
- T31S (p.Thr31Ser), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10022, NCI-TCGA Cosmic COSV5633, REVEL 0.01, CADD 8.26, Variant assessed as somatic; moderate impact.
- E32D (p.Glu32Asp), NCI-TCGA Cosmic COSV5634, MetaLR 0.02, MetaSVM -0.99, Variant assessed as somatic; moderate impact.
- E32V (p.Glu32Val), NCI-TCGA TCGA novel, REVEL 0.03, CADD 7.48, Variant assessed as somatic; moderate impact.
- S33* (p.Ser33Ter), rs2039690812, ClinGen CA344905026, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10023, CADD 35.00, Pathogenic
- S33P (p.Ser33Pro), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R34* (p.Arg34Ter), rs772808534, ClinGen CA1396855, cosmic curated COSV10813, ClinVar RCV000504668, CADD 35.00, Pathogenic
- R34Q (p.Arg34Gln), rs2039690682, ClinGen CA344905022, NCI-TCGA Cosmic COSV5637, cosmic curated COSV56373, REVEL 0.05, CADD 3.28, Uncertain significance
- G35C (p.Gly35Cys), TOPMed rs984551430, gnomAD rs984551430, REVEL 0.52, CADD 25.60
- G35R (p.Gly35Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L36F (p.Leu36Phe), NCI-TCGA Cosmic COSV5643, cosmic curated COSV56434, REVEL 0.04, CADD 18.60, Variant assessed as somatic; moderate impact.
- L36I (p.Leu36Ile), NCI-TCGA Cosmic COSV5643, Variant assessed as somatic; moderate impact.
- F37I (p.Phe37Ile), gnomAD rs1302813957, REVEL 0.43, CADD 25.50
- F37Y (p.Phe37Tyr), rs2039690517, ClinGen CA344905005, ClinVar RCV003013731, TOPMed rs2039690517, REVEL 0.32, CADD 25.30, Uncertain significance, not provided
- P38S (p.Pro38Ser), NCI-TCGA TCGA novel, REVEL 0.36, CADD 23.90, Variant assessed as somatic; moderate impact.
- P38T (p.Pro38Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R39G (p.Arg39Gly), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R39K (p.Arg39Lys), rs2102789073, ClinGen CA344904988, cosmic curated COSV10731, ClinVar RCV001905276, AlphaMissense 0.11, MetaLR 0.04, Uncertain significance, not provided
- R39M (p.Arg39Met), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10022, MetaLR 0.12, MetaSVM -1.00, Variant assessed as somatic; moderate impact.
- R39S (p.Arg39Ser), rs761822130, ClinGen CA1396853, ClinVar RCV002659543, ExAC rs761822130, REVEL 0.22, CADD 22.80, Uncertain significance, not provided
- E41A (p.Glu41Ala), TOPMed rs1211535189
- E41K (p.Glu41Lys), Ensembl rs2102789060
- E41V (p.Glu41Val), rs1211535189, ClinGen CA344904957, ClinVar RCV002801521, AlphaMissense 0.35, MetaLR 0.04, Uncertain significance, not provided
- N42K (p.Asn42Lys), rs774473277, ClinGen CA344904929, ClinVar RCV002272769, ExAC rs774473277, REVEL 0.27, CADD 3.00, Uncertain significance, Cone-rod dystrophy 3
- V43M (p.Val43Met), rs147421006, ClinGen CA1396851, ClinVar RCV001051408, ClinVar RCV001277093, REVEL 0.08, CADD 22.60, Uncertain significance
- G44E (p.Gly44Glu), rs2039690182, ClinGen CA344904907, cosmic curated COSV56452, ClinVar RCV001073479, REVEL 0.25, CADD 23.20, Uncertain significance, in USH2A
- G44R (p.Gly44Arg), rs1381795491, UniProt VAR 071996, gnomAD rs1381795491, REVEL 0.40, CADD 24.40, Pathogenic, in USH2A
- A45V (p.Ala45Val), TOPMed rs1025984020, MetaLR 0.15, MetaSVM -0.89
- F46Y (p.Phe46Tyr), rs2102789019, ClinGen CA344904879, cosmic curated COSV10813, ClinVar RCV001870902, REVEL 0.07, CADD 24.60, Uncertain significance, not provided
- K47N (p.Lys47Asn), NCI-TCGA Cosmic COSV5642, cosmic curated COSV56429, Uncertain significance, not provided
- K47Q (p.Lys47Gln), Ensembl rs2039690104, MetaLR 0.13, MetaSVM -0.78
- K48E (p.Lys48Glu), gnomAD rs1243255003, REVEL 0.02, CADD 17.60, Uncertain significance, Usher syndrome type 2A
- K48R (p.Lys48Arg), TOPMed rs2039690023, gnomAD rs2039690023, REVEL 0.03, CADD 12.00
- V49D (p.Val49Asp), rs1553258115, ClinGen CA344904824, ClinVar RCV000658551, Ensembl rs1553258115, AlphaMissense 0.53, MetaLR 0.14, Uncertain significance
- S50C (p.Ser50Cys), 1000Genomes rs200075564, REVEL 0.17, CADD 23.20
- S50F (p.Ser50Phe), cosmic curated COSV10513, 1000Genomes rs200075564, MetaLR 0.17, MetaSVM -0.90
- I51F (p.Ile51Phe), rs886043442, ClinGen CA344904800, ClinVar RCV001073546, TOPMed rs886043442, AlphaMissense 0.06, MetaLR 0.02, Uncertain significance
- I51V (p.Ile51Val), rs886043442, ClinGen CA10605529, ClinVar RCV000350826, TOPMed rs886043442, REVEL 0.01, AlphaMissense 0.06, Uncertain significance
- V52M (p.Val52Met), rs749099959, NCI-TCGA Cosmic COSV5632, cosmic curated COSV56322, ExAC rs749099959, REVEL 0.05, CADD 23.00, Variant assessed as somatic; moderate impact.
- P53A (p.Pro53Ala), rs2527655087, ClinGen CA344904773, ClinVar RCV003048180, Uncertain significance, not provided
- T54A (p.Thr54Ala), TOPMed rs2039689666, REVEL 0.08, CADD 0.97
- Q55* (p.Gln55Ter), rs2102788946, ClinGen CA344904733, ClinVar RCV001542517, Ensembl rs2102788946, Pathogenic
- A56S (p.Ala56Ser), NCI-TCGA TCGA novel, MetaLR 0.15, MetaSVM -0.94, Variant assessed as somatic; moderate impact.
- A56T (p.Ala56Thr), rs2102788940, ClinGen CA344904721, ClinVar RCV001922538, Ensembl rs2102788940, REVEL 0.23, CADD 23.60, Uncertain significance, not provided
- V57A (p.Val57Ala), Ensembl rs992877891, REVEL 0.04, CADD 9.84
- V57I (p.Val57Ile), NCI-TCGA TCGA novel, REVEL 0.04, CADD 9.04, Variant assessed as somatic; moderate impact.
- C58R (p.Cys58Arg), rs2039689429, ClinGen CA344904689, ClinVar RCV001928650, gnomAD rs2039689429, REVEL 0.47, CADD 24.00, Pathogenic, not provided
- C58Y (p.Cys58Tyr), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10023, MetaLR 0.21, MetaSVM -0.68, Uncertain significance, Usher syndrome type 2A
- G59E (p.Gly59Glu), rs1378799607, ClinGen CA344904669, ClinVar RCV001268038, ClinVar RCV003462845, REVEL 0.80, CADD 23.80, Likely pathogenic
- P61L (p.Pro61Leu), cosmic curated COSV10513, TOPMed rs938662688, gnomAD rs938662688, REVEL 0.13, CADD 22.70, Uncertain significance
- P61Q (p.Pro61Gln), rs938662688, ClinGen CA37922148, ClinVar RCV000601357, ClinVar RCV001829716, REVEL 0.08, CADD 18.50, Uncertain significance
- D62H (p.Asp62His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- D62N (p.Asp62Asn), rs567937233, ClinGen CA1396847, ClinVar RCV001058100, ClinVar RCV001099315, REVEL 0.01, CADD 3.12, Uncertain significance
- D62Y (p.Asp62Tyr), 1000Genomes rs567937233, ExAC rs567937233, TOPMed rs567937233, gnomAD rs567937233, REVEL 0.06, CADD 9.96, Uncertain significance
- R63* (p.Arg63Ter), rs781223647, ClinGen CA1396846, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10024, CADD 26.10, Pathogenic
- R63P (p.Arg63Pro), rs369806765, ClinGen CA344904640, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10024, REVEL 0.03, CADD 10.80, Uncertain significance
- R63Q (p.Arg63Gln), rs369806765, ClinGen CA1396845, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10453, REVEL 0.04, CADD 10.30, Uncertain significance
- S64N (p.Ser64Asn), rs778199517, ClinGen CA1396843, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10022, REVEL 0.03, CADD 16.60, Uncertain significance
- T65P (p.Thr65Pro), 1000Genomes rs200741942, ExAC rs200741942, gnomAD rs200741942, REVEL 0.06, CADD 14.50
- F66V (p.Phe66Val), NCI-TCGA Cosmic COSV5643, cosmic curated COSV56438, MetaLR 0.07, MetaSVM -0.96, Uncertain significance, Usher syndrome type 2A
- C67* (p.Cys67Ter), rs2527654883, ClinGen CA344904576, ClinVar RCV003696128, Pathogenic
- C67G (p.Cys67Gly), rs2102788868, ClinGen CA344904584, ClinVar RCV001787431, Ensembl rs2102788868, AlphaMissense 0.71, MetaLR 0.20, Likely pathogenic, Usher syndrome type 2A
- C67R (p.Cys67Arg), rs2102788868, ClinGen CA344904586, ClinVar RCV003890615, AlphaMissense 0.71, MetaLR 0.20, Likely pathogenic, Retinal dystrophy
- H68L (p.His68Leu), rs765666540, ClinGen CA37922147, NCI-TCGA Cosmic COSV1002, cosmic curated COSV10024, AlphaMissense 0.09, MetaLR 0.05, Uncertain significance, not provided
- H68P (p.His68Pro), ExAC rs765666540, gnomAD rs765666540, REVEL 0.07, AlphaMissense 0.09, Uncertain significance
- H68Y (p.His68Tyr), Ensembl rs1457417823, REVEL 0.04, CADD 17.80
- S69I (p.Ser69Ile), rs377254440, ClinGen CA1396838, ClinVar RCV000667934, ClinVar RCV001844213, REVEL 0.16, CADD 23.00, Uncertain significance
- S69N (p.Ser69Asn), ESP rs377254440, ExAC rs377254440, TOPMed rs377254440, gnomAD rs377254440, MetaLR 0.11, MetaSVM -0.77, Uncertain significance
- A71P (p.Ala71Pro), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10022, Variant assessed as somatic; moderate impact.
- A72G (p.Ala72Gly), TOPMed rs1320748695, gnomAD rs1320748695, REVEL 0.01, CADD 10.50
- A72T (p.Ala72Thr), ESP rs140476319, ExAC rs140476319
- A72V (p.Ala72Val), TOPMed rs1320748695, gnomAD rs1320748695, MetaLR 0.04, MetaSVM -1.01
- A73T (p.Ala73Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A73V (p.Ala73Val), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10023, MetaLR 0.04, MetaSVM -0.98, Variant assessed as somatic; moderate impact.
- E74A (p.Glu74Ala), rs774419989, ClinGen CA344904479, ClinVar RCV001230511, ExAC rs774419989, AlphaMissense 0.10, MetaLR 0.04, Uncertain significance
- E74G (p.Glu74Gly), ExAC rs774419989, TOPMed rs774419989, gnomAD rs774419989, REVEL 0.02, AlphaMissense 0.10, Uncertain significance
- E74K (p.Glu74Lys), cosmic curated COSV10453, TOPMed rs1342018128, gnomAD rs1342018128, REVEL 0.04, CADD 15.50
- S75N (p.Ser75Asn), rs768424417, ClinGen CA344904464, ClinVar RCV002720930, ExAC rs768424417, REVEL 0.07, CADD 13.30, Uncertain significance, not provided
- S75T (p.Ser75Thr), ExAC rs768424417, gnomAD rs768424417, REVEL 0.02, CADD 16.40, Uncertain significance
- Q77E (p.Gln77Glu), NCI-TCGA Cosmic COSV5634, cosmic curated COSV56347, Variant assessed as somatic; moderate impact.
- Q77L (p.Gln77Leu), NCI-TCGA Cosmic COSV5632, cosmic curated COSV56326, MetaLR 0.04, MetaSVM -0.99, Variant assessed as somatic; moderate impact.
- F78L (p.Phe78Leu), gnomAD rs1165607839, NCI-TCGA Cosmic COSV5632, cosmic curated COSV56326, REVEL 0.06, CADD 8.47, Variant assessed as somatic; moderate impact.
- F78V (p.Phe78Val), rs775094277, ClinGen CA1396832, ClinVar RCV000674232, ClinVar RCV001300495, REVEL 0.01, CADD 9.20, Pathogenic
- C79R (p.Cys79Arg), rs2527654698, ClinGen CA344904407, ClinVar RCV003066074, REVEL 0.56, CADD 24.60, Uncertain significance, not provided
- Q81K (p.Gln81Lys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R82G (p.Arg82Gly), ESP rs373005305, ExAC rs373005305, TOPMed rs373005305, gnomAD rs373005305, REVEL 0.10, CADD 15.60
- R82P (p.Arg82Pro), TOPMed rs1373263514, gnomAD rs1373263514, REVEL 0.15, CADD 21.20, Uncertain significance, Usher syndrome type 2A
- R82Q (p.Arg82Gln), cosmic curated COSV10453, TOPMed rs1373263514, gnomAD rs1373263514, REVEL 0.02, CADD 11.70
- R82W (p.Arg82Trp), ESP rs373005305, ExAC rs373005305, TOPMed rs373005305, gnomAD rs373005305, REVEL 0.14, CADD 21.90
- C84W (p.Cys84Trp), rs2039687530, ClinGen CA344904366, ClinVar RCV003239164, Uncertain significance, not provided
- C84Y (p.Cys84Tyr), rs1247310031, ClinGen CA344904369, ClinVar RCV001297295, Ensembl rs1247310031, AlphaMissense 0.90, MetaLR 0.20, Likely pathogenic
- I85F (p.Ile85Phe), rs770983063, ClinGen CA344904364, ClinVar RCV002644341, ExAC rs770983063, REVEL 0.07, CADD 3.04, Uncertain significance, not provided
- I85V (p.Ile85Val), rs770983063, ClinGen CA1396828, cosmic curated COSV56412, ClinVar RCV000512791, REVEL 0.03, CADD 0.00, Uncertain significance
- Q86E (p.Gln86Glu), NCI-TCGA Cosmic COSV5641, Variant assessed as somatic; moderate impact.
- Q86K (p.Gln86Lys), NCI-TCGA Cosmic COSV5641, cosmic curated COSV56410, Variant assessed as somatic; moderate impact.
- Q86L (p.Gln86Leu), rs747033392, ClinGen CA344904354, ClinVar RCV003881686, AlphaMissense 0.15, MetaLR 0.14, Uncertain significance, Usher syndrome type 2A
- Q86R (p.Gln86Arg), cosmic curated COSV56374, ExAC rs747033392, gnomAD rs747033392, REVEL 0.24, AlphaMissense 0.15
- C88* (p.Cys88Ter), rs368798834, ClinGen CA344904337, ClinVar RCV001093205, ClinVar RCV005633886, CADD 26.20, Pathogenic
- C88F (p.Cys88Phe), rs2039687321, ClinGen CA344904338, NCI-TCGA Cosmic COSV5638, cosmic curated COSV56385, AlphaMissense 0.74, MetaLR 0.21, Uncertain significance
- C88S (p.Cys88Ser), rs2102788720, ClinGen CA344904343, ClinVar RCV001929986, Ensembl rs2102788720, AlphaMissense 0.87, MetaLR 0.20, Likely pathogenic, not provided
- C88W (p.Cys88Trp), rs368798834, ClinGen CA143444, ClinVar RCV000041815, ClinVar RCV000666896, REVEL 0.36, CADD 16.90, Pathogenic
- P89A (p.Pro89Ala), ExAC rs758792895, TOPMed rs758792895, gnomAD rs758792895, REVEL 0.46, CADD 23.70, Uncertain significance
- P89L (p.Pro89Leu), ExAC rs753270541, gnomAD rs753270541, REVEL 0.46, CADD 24.30
- P89S (p.Pro89Ser), rs758792895, ClinGen CA1396826, ClinVar RCV004484432, ClinVar RCV004759398, REVEL 0.40, CADD 24.20, Uncertain significance, Inborn genetic diseases; not provided
- Y90C (p.Tyr90Cys), rs755435330, ClinGen CA1396823, ClinVar RCV001953352, ClinVar RCV003475194, REVEL 0.65, CADD 22.80, Pathogenic/Likely pathogenic, Retinitis pigmentosa 39; not provided
- Y90H (p.Tyr90His), ExAC rs779127191, gnomAD rs779127191, REVEL 0.02, CADD 5.48
- R91* (p.Arg91Ter), rs2527654487, ClinGen CA344904325, ClinVar RCV003682548, Pathogenic
- R91I (p.Arg91Ile), NCI-TCGA Cosmic COSV1002, Variant assessed as somatic; moderate impact.
- R91K (p.Arg91Lys), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10023, MetaLR 0.08, MetaSVM -0.94, Variant assessed as somatic; moderate impact.
- S92A (p.Ser92Ala), rs192918169, ClinGen CA1396822, ClinVar RCV001733053, ClinVar RCV003451865, REVEL 0.10, CADD 22.90, Uncertain significance, Retinitis pigmentosa 39; Inborn genetic diseases; Usher syndrome type 2A
- H94Q (p.His94Gln), TOPMed rs1231616703, gnomAD rs1231616703, REVEL 0.03, CADD 5.91, Uncertain significance, Inborn genetic diseases
- P95H (p.Pro95His), cosmic curated COSV10024, Ensembl rs1283365398, MetaLR 0.18, MetaSVM -0.88
- P95T (p.Pro95Thr), rs767339477, ClinGen CA1396821, ClinVar RCV003118557, ExAC rs767339477, REVEL 0.04, CADD 14.90, Uncertain significance, not provided
- T96A (p.Thr96Ala), rs557642490, ClinGen CA1396820, ClinVar RCV001364475, ClinVar RCV001826031, REVEL 0.01, CADD 0.00, Uncertain significance
- T96I (p.Thr96Ile), Ensembl rs2039686699, MetaLR 0.03, MetaSVM -1.03
- T96P (p.Thr96Pro), ExAC rs557642490, TOPMed rs557642490, gnomAD rs557642490, REVEL 0.01, CADD 0.00, Uncertain significance
- T98A (p.Thr98Ala), TOPMed rs2039686492, gnomAD rs2039686492, REVEL 0.02, CADD 0.06
- T98S (p.Thr98Ser), NCI-TCGA Cosmic COSV5642, cosmic curated COSV56424, MetaLR 0.03, MetaSVM -1.01, Variant assessed as somatic; moderate impact.
- A99S (p.Ala99Ser), NCI-TCGA TCGA novel, REVEL 0.03, CADD 4.52, Variant assessed as somatic; moderate impact.
- A99T (p.Ala99Thr), rs2039686454, ClinGen CA344904276, ClinVar RCV001229536, Ensembl rs2039686454, AlphaMissense 0.09, MetaLR 0.04, Uncertain significance
- A99V (p.Ala99Val), NCI-TCGA Cosmic COSV5636, cosmic curated COSV56362, REVEL 0.02, CADD 7.36, Variant assessed as somatic; moderate impact.
- L100F (p.Leu100Phe), rs1425614240, NCI-TCGA Cosmic COSV5639, cosmic curated COSV56391, TOPMed rs1425614240, REVEL 0.13, CADD 23.70, Variant assessed as somatic; moderate impact.
- L100H (p.Leu100His), rs1558082163, ClinGen CA344904267, ClinVar RCV001073705, Ensembl rs1558082163, AlphaMissense 0.33, MetaLR 0.18, Uncertain significance
- L100P (p.Leu100Pro), rs1558082163, ClinGen CA344904266, ClinVar RCV000733244, Ensembl rs1558082163, REVEL 0.30, AlphaMissense 0.33, Uncertain significance
- F101L (p.Phe101Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- F101S (p.Phe101Ser), Ensembl rs2039686229, MetaLR 0.08, MetaSVM -1.07
- S102* (p.Ser102Ter), NCI-TCGA Cosmic COSV1002, cosmic curated COSV10023, Variant assessed as somatic; high impact.
Public USH2A analysis runs
- USH2A analysis run — USH2A (8,895 variants) — completed 2026-08-19