SPTBN2 (O15020) variants and mutations
SPTBN2 (also known as O15020) is a human protein-coding gene encoding a spectrin beta chain, non-erythrocytic 2 protein. It organizes the neuronal membrane cytoskeleton and is particularly important for Purkinje-cell structure and signaling in the cerebellum. Dominant variants cause spinocerebellar ataxia type 5 or early-onset developmental ataxia, while biallelic variants can cause a more severe SCAR phenotype. This analysis covers 3,169 SPTBN2 variants and mutations. Of these, 70% have computational variant effect predictions. Disease context includes spinocerebellar ataxia type 5, autosomal recessive spinocerebellar ataxia 14, and Spectrin-associated autosomal recessive cerebellar ataxia. Example SPTBN2 variants include S2R, T4A, and T4K.
Variant analysis overview
- Gene: SPTBN2
- Protein: O15020
- UniProt accession: O15020
- Organism: Homo sapiens
- Variants analyzed: 3169
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 2,897 unspecified-consequence records; 8 in-frame deletions; 91 synonymous variants; 145 missense variants; 5 stop-gained variants; 15 frameshift variants; 2 splice-region variants; 1 stop retained variant; 1 in-frame insertions; 4 substitution
- Prediction scores: 2,223 variants have prediction scores (70% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: spinocerebellar ataxia type 5, autosomal recessive spinocerebellar ataxia 14, Spectrin-associated autosomal recessive cerebellar ataxia, hereditary disease, cerebellar ataxia, spinocerebellar ataxia type 14, Intellectual disability, stroke disorder, alcohol drinking, hereditary ataxia, hereditary spastic paraplegia, genetic developmental and epileptic encephalopathy.
Protein structure and variant hotspots
- Protein features: 3 domains; 9 post-translational modification sites.
- Structural context: 458 variants have structural context.
- PTM context: 11 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable SPTBN2 variants
Examples include S2R, T4A, T4K, T4M, S6L, S6T, P7L, T8A. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- S2R (p.Ser2Arg), cosmic curated COSV59459
- T4A (p.Thr4Ala), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- T4K (p.Thr4Lys), rs749463565, ClinGen CA224101734, ClinVar RCV003553610, ClinVar RCV004731545, REVEL 0.23, CADD 22.90, Uncertain significance, not provided; Inborn genetic diseases
- T4M (p.Thr4Met), rs749463565, NCI-TCGA Cosmic COSV1000, cosmic curated COSV10002, ExAC rs749463565, REVEL 0.26, CADD 19.50, Uncertain significance
- S6L (p.Ser6Leu), NCI-TCGA Cosmic COSV5946, cosmic curated COSV59460, TOPMed rs1942386577, REVEL 0.32, CADD 24.20, Variant assessed as somatic; moderate impact.
- S6T (p.Ser6Thr), TOPMed rs1942386777, REVEL 0.25, CADD 23.20
- P7L (p.Pro7Leu), TOPMed rs1239445065, REVEL 0.16, CADD 23.20
- T8A (p.Thr8Ala), ExAC rs773027732, TOPMed rs773027732, gnomAD rs773027732, REVEL 0.17, CADD 21.60
- T8R (p.Thr8Arg), gnomAD rs1235974980, REVEL 0.21, CADD 25.30
- F10V (p.Phe10Val), NCI-TCGA TCGA novel, REVEL 0.17, CADD 22.60, Variant assessed as somatic; moderate impact.
- S12R (p.Ser12Arg), cosmic curated COSV59458, REVEL 0.28, CADD 24.80
- Q16H (p.Gln16His), ExAC rs747934235, gnomAD rs747934235
- Q18H (p.Gln18His), rs377573278, ClinGen CA6129780, ClinVar RCV002999464, ClinVar RCV004963340, REVEL 0.15, CADD 24.30, Conflicting interpretations, not provided; Inborn genetic diseases
- S20G (p.Ser20Gly), ExAC rs781276338, gnomAD rs781276338, REVEL 0.15, CADD 24.70
- S20N (p.Ser20Asn), TOPMed rs1023961480, Uncertain significance, Inborn genetic diseases
- D21N (p.Asp21Asn), TOPMed rs1942384174
- D21Y (p.Asp21Tyr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- N23S (p.Asn23Ser), Ensembl rs2135559335
- R25C (p.Arg25Cys), TOPMed rs1399781384, REVEL 0.51, CADD 32.00
- R25L (p.Arg25Leu), gnomAD rs1942383868, REVEL 0.33, CADD 25.50
- W26* (p.Trp26Ter), cosmic curated COSV10462, Ensembl rs1565157355
- D27N (p.Asp27Asn), TOPMed rs1013903563
- L28F (p.Leu28Phe), rs2496681462, ClinGen CA381485216, ClinVar RCV002797137, Uncertain significance, not provided
- P29L (p.Pro29Leu), rs1257151945, NCI-TCGA Cosmic COSV5944, cosmic curated COSV59445, gnomAD rs1257151945, REVEL 0.10, CADD 22.80, Variant assessed as somatic; moderate impact.
- P29T (p.Pro29Thr), TOPMed rs1942383524, gnomAD rs1942383524, REVEL 0.04, CADD 21.50
- S31L (p.Ser31Leu), rs147766428, ClinGen CA6129776, ClinVar RCV000585022, ClinVar RCV002244994, REVEL 0.07, CADD 22.30, Conflicting interpretations, Inborn genetic diseases; Autosomal recessive spinocerebellar ataxia 14; Spinocer
- S31P (p.Ser31Pro), rs373669452, ClinGen CA6129777, ClinVar RCV000500765, ESP rs373669452, REVEL 0.12, CADD 21.80, Uncertain significance, not specified
- D32E (p.Asp32Glu), TOPMed rs1942382845, REVEL 0.06, CADD 13.60
- D32Y (p.Asp32Tyr), rs935849810, ClinGen CA224101627, ClinVar RCV002892600, TOPMed rs935849810, REVEL 0.28, CADD 25.90, Uncertain significance, Inborn genetic diseases
- N35I (p.Asn35Ile), ESP rs370531619, ExAC rs370531619, TOPMed rs370531619, gnomAD rs370531619, REVEL 0.26, CADD 26.20
- N35S (p.Asn35Ser), ESP rs370531619, ExAC rs370531619, TOPMed rs370531619, gnomAD rs370531619, REVEL 0.12, CADD 21.80
- D36G (p.Asp36Gly), ExAC rs765521246, gnomAD rs765521246, REVEL 0.11, CADD 22.60
- D36V (p.Asp36Val), ExAC rs765521246, gnomAD rs765521246
- S37G (p.Ser37Gly), ExAC rs760026876, gnomAD rs760026876, REVEL 0.08, CADD 23.70
- S37R (p.Ser37Arg), cosmic curated COSV10811
- S39L (p.Ser39Leu), NCI-TCGA TCGA novel, REVEL 0.33, CADD 28.50, Variant assessed as somatic; moderate impact.
- A40V (p.Ala40Val), cosmic curated COSV10001, Uncertain significance, not specified
- R41C (p.Arg41Cys), rs1942382097, ClinGen CA381485068, ClinVar RCV002927017, TOPMed rs1942382097, REVEL 0.35, CADD 26.80, Uncertain significance, not provided
- R41H (p.Arg41His), rs149103293, ClinGen CA6129766, cosmic curated COSV10964, ClinVar RCV002581372, REVEL 0.31, CADD 26.40, Conflicting interpretations, not provided; Inborn genetic diseases
- R41L (p.Arg41Leu), cosmic curated COSV10882, 1000Genomes rs149103293, ESP rs149103293, ExAC rs149103293, REVEL 0.34, CADD 26.30, Likely benign
- E44Q (p.Glu44Gln), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S46A (p.Ser46Ala), Ensembl rs1590981699
- R47C (p.Arg47Cys), rs1378267921, ClinGen CA381484994, ClinVar RCV002882808, TOPMed rs1378267921, REVEL 0.41, CADD 26.10, Uncertain significance, Inborn genetic diseases
- R47H (p.Arg47His), rs768391963, NCI-TCGA Cosmic COSV1000, cosmic curated COSV10002, ExAC rs768391963, REVEL 0.37, CADD 26.80, Variant assessed as somatic; moderate impact.
- R47L (p.Arg47Leu), ExAC rs768391963, gnomAD rs768391963, REVEL 0.56, CADD 26.40
- I48V (p.Ile48Val), TOPMed rs1198850466
- K49E (p.Lys49Glu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- K49N (p.Lys49Asn), NCI-TCGA Cosmic COSV5944, cosmic curated COSV59449, Variant assessed as somatic; moderate impact.
- A50V (p.Ala50Val), cosmic curated COSV10590
- L51V (p.Leu51Val), gnomAD rs1439956051, REVEL 0.27, CADD 23.40
- D53G (p.Asp53Gly), gnomAD rs1942127203, REVEL 0.49, CADD 29.30
- D53Y (p.Asp53Tyr), cosmic curated COSV10001
- E54Q (p.Glu54Gln), TOPMed rs1942127067
- R55* (p.Arg55Ter), cosmic curated COSV10964, CADD 36.00
- R55Q (p.Arg55Gln), cosmic curated COSV59458, gnomAD rs1217789386, REVEL 0.47, CADD 27.00
- A57P (p.Ala57Pro), cosmic curated COSV59448
- V58L (p.Val58Leu), cosmic curated COSV59447
- V58M (p.Val58Met), rs1554989512, ClinGen CA381484419, cosmic curated COSV59451, ClinVar RCV000499933, Uncertain significance, not specified
- K61E (p.Lys61Glu), rs797046006, ClinGen CA205211, ClinVar RCV000192407, ClinVar RCV000494630, Likely pathogenic, Cerebellar ataxia; not provided
- K61N (p.Lys61Asn), rs2496577708, ClinVar RCV004575934, Uncertain significance, not provided
- T62I (p.Thr62Ile), rs2135526299, ClinGen CA381484385, ClinVar RCV003884003, Uncertain significance, Spinocerebellar ataxia type 5
- T62N (p.Thr62Asn), rs2135526299, ClinGen CA381484386, ClinVar RCV001994920, Ensembl rs2135526299, Conflicting interpretations, not provided
- F63L (p.Phe63Leu), rs2135526260, ClinGen CA381484377, ClinVar RCV002265088, Ensembl rs2135526260, Uncertain significance, not provided
- T64A (p.Thr64Ala), rs769557138, ClinGen CA6129743, ClinVar RCV001354818, ExAC rs769557138, REVEL 0.97, CADD 26.40, Uncertain significance, not provided
- K65Q (p.Lys65Gln), rs2135526204, ClinGen CA381484369, ClinVar RCV002221400, Ensembl rs2135526204, Likely pathogenic, Spinocerebellar ataxia type 5
- W66C (p.Trp66Cys), cosmic curated COSV10001
- V67I (p.Val67Ile), Ensembl rs1565151628
- S69L (p.Ser69Leu), cosmic curated COSV10518, ExAC rs773270398, gnomAD rs773270398, REVEL 0.89, CADD 28.00
- H70P (p.His70Pro), Ensembl rs1590970853
- L71P (p.Leu71Pro), gnomAD rs1241364345, REVEL 0.92, CADD 28.70
- A72S (p.Ala72Ser), NCI-TCGA Cosmic COSV1000, cosmic curated COSV10002, Variant assessed as somatic; moderate impact.
- A72T (p.Ala72Thr), cosmic curated COSV10001
- R73G (p.Arg73Gly), ExAC rs536375005, TOPMed rs536375005, gnomAD rs536375005
- R73Q (p.Arg73Gln), gnomAD rs1300028290, REVEL 0.27, CADD 26.20, Uncertain significance, Inborn genetic diseases
- R73W (p.Arg73Trp), rs536375005, NCI-TCGA Cosmic COSV5945, cosmic curated COSV59459, ExAC rs536375005, REVEL 0.59, CADD 28.90, Uncertain significance, Inborn genetic diseases
- T75M (p.Thr75Met), rs369925402, ClinGen CA6129737, cosmic curated COSV59454, ClinVar RCV003816474, REVEL 0.40, CADD 27.30, Uncertain significance, not provided
- C76G (p.Cys76Gly), ExAC rs780472257, gnomAD rs780472257, REVEL 0.52, CADD 26.80
- C76R (p.Cys76Arg), ExAC rs780472257, gnomAD rs780472257, REVEL 0.58, CADD 26.80
- R77G (p.Arg77Gly), rs200956071, ClinVar RCV004592418, Uncertain significance, not provided
- R77Q (p.Arg77Gln), cosmic curated COSV10518, 1000Genomes rs183081994, ExAC rs183081994, gnomAD rs183081994, REVEL 0.40, CADD 26.70, Uncertain significance, not provided
- R77W (p.Arg77Trp), rs200956071, ClinGen CA243402, ClinVar RCV000177266, ClinVar RCV003278678, REVEL 0.47, CADD 29.60, Conflicting interpretations, Inborn genetic diseases; not provided
- V78L (p.Val78Leu), ESP rs149918123, ExAC rs149918123, TOPMed rs149918123, gnomAD rs149918123, Uncertain significance
- V78M (p.Val78Met), rs149918123, ClinGen CA6129732, ClinVar RCV001289191, ESP rs149918123, REVEL 0.73, CADD 25.20, Uncertain significance, Inborn genetic diseases; not provided
- G79A (p.Gly79Ala), TOPMed rs1942122301, REVEL 0.13, CADD 16.40, Uncertain significance, Inborn genetic diseases
- D80E (p.Asp80Glu), ExAC rs775075817, gnomAD rs775075817
- D80N (p.Asp80Asn), ExAC rs762677201, TOPMed rs762677201, gnomAD rs762677201, REVEL 0.43, CADD 26.60
- D80Y (p.Asp80Tyr), cosmic curated COSV59448
- L81M (p.Leu81Met), cosmic curated COSV10002, Ensembl rs772427786, REVEL 0.77, CADD 24.60
- Y82C (p.Tyr82Cys), NCI-TCGA Cosmic COSV5944, cosmic curated COSV59446, REVEL 0.76, CADD 28.50, Variant assessed as somatic; moderate impact.
- S83G (p.Ser83Gly), rs765078549, ClinGen CA6129727, ClinVar RCV004457921, ExAC rs765078549, REVEL 0.28, CADD 22.10, Uncertain significance, Inborn genetic diseases
- D84N (p.Asp84Asn), cosmic curated COSV59446, gnomAD rs1272630539, REVEL 0.80, CADD 26.20
- L85H (p.Leu85His), cosmic curated COSV10964
- L85P (p.Leu85Pro), rs2496574851, ClinGen CA381484241, ClinVar RCV003338158, Uncertain significance, Autosomal recessive spinocerebellar ataxia 14
- R86Q (p.Arg86Gln), ExAC rs770888940, TOPMed rs770888940, gnomAD rs770888940, REVEL 0.36, CADD 26.70
- R86W (p.Arg86Trp), rs776593274, NCI-TCGA Cosmic COSV5945, cosmic curated COSV59451, ExAC rs776593274, REVEL 0.73, CADD 27.90, Variant assessed as somatic; moderate impact.
- G88L (p.Gly88Leu), cosmic curated COSV59453
- R89C (p.Arg89Cys), rs1565151375, ClinGen CA381484210, cosmic curated COSV59449, ClinVar RCV000713036, REVEL 0.40, CADD 26.70, Uncertain significance, not provided
- R89H (p.Arg89His), rs374485184, ClinGen CA6129721, NCI-TCGA Cosmic COSV5944, cosmic curated COSV59446, REVEL 0.38, CADD 25.70, Uncertain significance, not specified; not provided; Inborn genetic diseases
- R89L (p.Arg89Leu), rs374485184, ClinGen CA6129722, ClinVar RCV003482022, ClinVar RCV005744681, REVEL 0.36, CADD 25.40, Uncertain significance, Inborn genetic diseases; not provided
- R89P (p.Arg89Pro), cosmic curated COSV59462
- R89S (p.Arg89Ser), cosmic curated COSV59463
- N90S (p.Asn90Ser), ExAC rs749591934, TOPMed rs749591934, gnomAD rs749591934, REVEL 0.35, CADD 22.40
- R93S (p.Arg93Ser), 1000Genomes rs191736279, ExAC rs191736279, TOPMed rs191736279, gnomAD rs191736279, REVEL 0.35, CADD 18.80
- L94F (p.Leu94Phe), rs2496573714, ClinGen CA381484162, ClinVar RCV004457922, Uncertain significance, Inborn genetic diseases
- L95F (p.Leu95Phe), NCI-TCGA Cosmic COSV5946, cosmic curated COSV59462, Variant assessed as somatic; moderate impact.
- E96K (p.Glu96Lys), Ensembl rs986153925, REVEL 0.78, CADD 25.30
- V97G (p.Val97Gly), Ensembl rs1590970534
- V97M (p.Val97Met), TOPMed rs1401862278, gnomAD rs1401862278, REVEL 0.45, CADD 24.10
- L98F (p.Leu98Phe), cosmic curated COSV59460
- S99L (p.Ser99Leu), cosmic curated COSV10002, TOPMed rs1171949662, gnomAD rs1171949662, REVEL 0.95, CADD 25.90
- E101D (p.Glu101Asp), Ensembl rs2135525263
- I102Y (p.Ile102Tyr), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- L103=, NCI-TCGA TCGA novel, Variant assessed as somatic; low impact.
- P104S (p.Pro104Ser), gnomAD rs1942089761, REVEL 0.71, CADD 33.00
- P106H (p.Pro106His), cosmic curated COSV59462
- K108N (p.Lys108Asn), ESP rs143691410, ExAC rs143691410, TOPMed rs143691410, gnomAD rs143691410, REVEL 0.47, CADD 24.30, Uncertain significance, not provided
- R110C (p.Arg110Cys), cosmic curated COSV59450, TOPMed rs1237726892, gnomAD rs1237726892, REVEL 0.56, CADD 30.00
- R110H (p.Arg110His), cosmic curated COSV10964, ExAC rs778491140, gnomAD rs778491140, REVEL 0.37, CADD 29.20
- R110S (p.Arg110Ser), cosmic curated COSV10002
- R112W (p.Arg112Trp), rs1309547051, NCI-TCGA Cosmic COSV5944, cosmic curated COSV59449, gnomAD rs1309547051, REVEL 0.72, CADD 25.90, Variant assessed as somatic; moderate impact.
- C115S (p.Cys115Ser), TOPMed rs1942088325, gnomAD rs1942088325, REVEL 0.45, CADD 24.20
- E117G (p.Glu117Gly), gnomAD rs1942088032, REVEL 0.63, CADD 33.00
- N118S (p.Asn118Ser), NCI-TCGA Cosmic COSV5945, cosmic curated COSV59458, Variant assessed as somatic; moderate impact.
- V119A (p.Val119Ala), Ensembl rs1942087617
- V119M (p.Val119Met), cosmic curated COSV10964, ExAC rs760516394, gnomAD rs760516394, REVEL 0.46, CADD 25.80
- D120N (p.Asp120Asn), Ensembl rs1565150741
- K121Q (p.Lys121Gln), 1000Genomes rs200462640, ExAC rs200462640, gnomAD rs200462640, REVEL 0.79, CADD 26.70
- K121R (p.Lys121Arg), ExAC rs764048472, gnomAD rs764048472, REVEL 0.71, CADD 27.60
- A122T (p.Ala122Thr), rs376084729, cosmic curated COSV59451, ESP rs376084729, ExAC rs376084729, Variant assessed as somatic; moderate impact.
- Q124R (p.Gln124Arg), gnomAD rs1164430196, REVEL 0.45, CADD 26.10
- L126F (p.Leu126Phe), cosmic curated COSV59462
- L126I (p.Leu126Ile), NCI-TCGA Cosmic COSV5946, Variant assessed as somatic; moderate impact.
- K127T (p.Lys127Thr), ESP rs140092196, ExAC rs140092196, TOPMed rs140092196, gnomAD rs140092196, REVEL 0.35, CADD 25.30
- E128* (p.Glu128Ter), ExAC rs777128229, TOPMed rs777128229, gnomAD rs777128229, CADD 36.00
- E128K (p.Glu128Lys), ExAC rs777128229, TOPMed rs777128229, gnomAD rs777128229, REVEL 0.63, CADD 26.90
- M136V (p.Met136Val), rs150610657, ClinGen CA6129677, ClinVar RCV000520202, ESP rs150610657, REVEL 0.32, CADD 22.50, Conflicting interpretations, not provided
- S138F (p.Ser138Phe), cosmic curated COSV59445, REVEL 0.68, CADD 28.60
- H139Y (p.His139Tyr), ExAC rs772480880, gnomAD rs772480880, REVEL 0.88, CADD 26.40
- D140N (p.Asp140Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- D140Y (p.Asp140Tyr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- I141S (p.Ile141Ser), TOPMed rs1942084458
- I141T (p.Ile141Thr), TOPMed rs1942084458
- G144R (p.Gly144Arg), rs2496554180, ClinGen CA381483660, ClinVar RCV002618384, REVEL 0.76, CADD 26.30, Uncertain significance, not provided
- R147* (p.Arg147Ter), TOPMed rs1817109370, CADD 36.00
- G151E (p.Gly151Glu), cosmic curated COSV59452
- V153I (p.Val153Ile), TOPMed rs1554989084, Uncertain significance
- V153L (p.Val153Leu), rs1554989084, ClinGen CA381483603, ClinVar RCV000517473, TOPMed rs1554989084, Uncertain significance, not specified
- W154L (p.Trp154Leu), cosmic curated COSV10001
- I156M (p.Ile156Met), ExAC rs779801896
- I156V (p.Ile156Val), ExAC rs753547565, TOPMed rs753547565, gnomAD rs753547565, REVEL 0.43, CADD 26.10, Uncertain significance, not provided
- I157F (p.Ile157Phe), rs2135521053, ClinGen CA381483577, ClinVar RCV002265437, Ensembl rs2135521053, Uncertain significance, not provided
- I157T (p.Ile157Thr), rs875989881, ClinGen CA10576252, ClinVar RCV000211499, Ensembl rs875989881, Likely pathogenic, Spinocerebellar ataxia type 5
- L158F (p.Leu158Phe), cosmic curated COSV10462
- R159* (p.Arg159Ter), cosmic curated COSV59450, ExAC rs755976699, TOPMed rs755976699, gnomAD rs755976699, CADD 37.00
- R159G (p.Arg159Gly), ExAC rs755976699, TOPMed rs755976699, gnomAD rs755976699, REVEL 0.77, CADD 27.60
- R159Q (p.Arg159Gln), rs886048552, ClinGen CA10639135, NCI-TCGA Cosmic COSV5944, cosmic curated COSV59449, REVEL 0.67, CADD 29.30, Uncertain significance, Inborn genetic diseases
- F160L (p.Phe160Leu), rs2496552835, ClinGen CA381483563, ClinVar RCV002290389, Uncertain significance, Spinocerebellar ataxia type 5
- F160S (p.Phe160Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- Q161H (p.Gln161His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S166R (p.Ser166Arg), TOPMed rs1942039262
- T169I (p.Thr169Ile), cosmic curated COSV59453
- E170K (p.Glu170Lys), TOPMed rs1942039120
- D171H (p.Asp171His), ExAC rs755741689, gnomAD rs755741689, REVEL 0.46, CADD 27.20
- D171N (p.Asp171Asn), ExAC rs755741689, gnomAD rs755741689, REVEL 0.29, CADD 27.70
- N172K (p.Asn172Lys), gnomAD rs1197833233, REVEL 0.10, CADD 21.50
- N172Y (p.Asn172Tyr), TOPMed rs1373599834, gnomAD rs1373599834, REVEL 0.29, CADD 25.60
- E174D (p.Glu174Asp), cosmic curated COSV10440
- E174K (p.Glu174Lys), NCI-TCGA Cosmic COSV1000, cosmic curated COSV10001, Variant assessed as somatic; moderate impact.
- K175* (p.Lys175Ter), gnomAD rs1431236793, CADD 37.00
- K175E (p.Lys175Glu), rs1431236793, ClinGen CA381483438, ClinVar RCV003329814, Uncertain significance, not provided
- K175R (p.Lys175Arg), gnomAD rs1269016964, REVEL 0.15, CADD 25.40, Uncertain significance, Inborn genetic diseases
- S177A (p.Ser177Ala), rs2496528994, ClinGen CA381483421, ClinVar RCV003277651, Uncertain significance, Inborn genetic diseases
- A178S (p.Ala178Ser), gnomAD rs1057524761, REVEL 0.42, CADD 24.80, Likely pathogenic
- A178T (p.Ala178Thr), rs1057524761, ClinGen CA16606980, ClinVar RCV000423934, gnomAD rs1057524761, Likely pathogenic, not provided
- A181T (p.Ala181Thr), rs2496528788, ClinGen CA381483396, ClinVar RCV003326837, Uncertain significance, not provided
- L183F (p.Leu183Phe), TOPMed rs1942037567, REVEL 0.84, CADD 25.80
- L184R (p.Leu184Arg), ExAC rs751600453, gnomAD rs751600453, REVEL 0.87, CADD 27.20
- W185* (p.Trp185Ter), Ensembl rs1565149618
- W185C (p.Trp185Cys), Ensembl rs1565149610
- W185L (p.Trp185Leu), cosmic curated COSV10605
Public SPTBN2 analysis runs
- SPTBN2 analysis run — SPTBN2 (3,169 variants) — completed 2026-08-19