SGCA (Alpha-sarcoglycan) variants and mutations
SGCA (also known as Alpha-sarcoglycan) is a human protein-coding gene encoding an alpha-sarcoglycan protein. It is part of the sarcoglycan complex that stabilizes the muscle-cell membrane during contraction by linking dystrophin-associated structures to extracellular matrix. Biallelic loss-of-function variants cause limb-girdle muscular dystrophy R3 with progressive proximal weakness and possible cardiomyopathy. This analysis covers 684 SGCA variants and mutations. Of these, 82% have computational variant effect predictions. Disease context includes autosomal recessive limb-girdle muscular dystrophy type 2D, autosomal recessive limb-girdle muscular dystrophy, and Abnormality of the musculature. Example SGCA variants include M1V, T4K, and T4T.
Variant analysis overview
- Gene: SGCA
- Protein: Alpha-sarcoglycan
- UniProt accession: Q16586
- Organism: Homo sapiens
- Variants analyzed: 684
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 549 unspecified-consequence records; 12 frameshift variants; 66 synonymous variants; 45 missense variants; 3 splice-region variants; 2 in-frame deletions; 3 stop-gained variants; 1 protein altering variant; 3 substitution
- Prediction scores: 558 variants have prediction scores (82% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: autosomal recessive limb-girdle muscular dystrophy type 2D, autosomal recessive limb-girdle muscular dystrophy, Abnormality of the musculature, sarcoglycanopathy, limb-girdle muscular dystrophy, muscular dystrophy, hereditary disease, Elevated circulating creatine kinase concentration, Alzheimer disease, qualitative or quantitative defects of alpha-sarcoglycan, Proximal muscle weakness, Thomsen and Becker disease.
Protein structure and variant hotspots
- Protein features: 1 transmembrane segments; 3 post-translational modification sites.
- Structural context: 18 variants have structural context.
- PTM context: 3 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable SGCA variants
Examples include M1V, T4K, T4T, L5V, F6L, F6I, F6F, W7*. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1V (p.Met1Val), rs2509113878, ClinGen CA400210471, ClinVar RCV002281872, ClinVar RCV003621621, Pathogenic/Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy; Autosomal recessive limb-gir
- T4K (p.Thr4Lys), NCI-TCGA Cosmic COSV5624, cosmic curated COSV56248, Variant assessed as somatic; moderate impact.
- T4T (p.Thr4Thr), gnomAD 17-50166052-A-G, CADD 0.90
- L5V (p.Leu5Val), rs2144488329, ClinGen CA400210586, ClinVar RCV001981335, Ensembl rs2144488329, REVEL 0.09, CADD 0.79, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- F6L (p.Phe6Leu), rs1189219411, gnomAD 17-50166049-GAC-G, CADD 15.30
- F6I (p.Phe6Ile), gnomAD 17-50166056-T-A, REVEL 0.19, CADD 0.04
- F6F (p.Phe6Phe), rs2144488335, gnomAD 17-50166058-C-T, CADD 12.90
- W7* (p.Trp7Ter), rs2509113935, ClinGen CA400210641, ClinVar RCV003472672, Likely pathogenic
- W7G (p.Trp7Gly), ExAC rs749990267, gnomAD rs749990267, REVEL 0.65, CADD 25.30
- W7F (p.Trp7Phe), gnomAD 17-50166055-C-CTT, CADD 9.85
- W7C (p.Trp7Cys), gnomAD 17-50166061-G-C, REVEL 0.69, CADD 28.30
- T8T (p.Thr8Thr), rs1165668797, gnomAD 17-50166064-T-A, CADD 2.60
- P9H (p.Pro9His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P9L (p.Pro9Leu), gnomAD rs1460300052, REVEL 0.17, CADD 1.18
- P9Q (p.Pro9Gln), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- P9T (p.Pro9Thr), gnomAD rs1420118468, REVEL 0.16, CADD 2.90
- P9P (p.Pro9Pro), gnomAD 17-50166067-T-C, CADD 10.40
- L10F (p.Leu10Phe), rs1904771955, ClinGen CA400210713, ClinVar RCV002633695, gnomAD rs1904771955, REVEL 0.31, CADD 7.75, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- L10R (p.Leu10Arg), rs2509113948, ClinGen CA2739268211, ClinVar RCV003622754, Pathogenic
- L10P (p.Leu10Pro), gnomAD 17-50166065-CCT-C, CADD 21.90
- L11F (p.Leu11Phe), rs1164863952, NCI-TCGA Cosmic COSV5625, cosmic curated COSV56251, TOPMed rs1164863952, REVEL 0.49, CADD 15.80, Variant assessed as somatic; moderate impact.
- L11L (p.Leu11Leu), rs762704751, gnomAD 17-50166073-C-T, CADD 8.21
- V12L (p.Val12Leu), ExAC rs766209304, TOPMed rs766209304, gnomAD rs766209304, REVEL 0.33, CADD 2.90, Uncertain significance
- V12M (p.Val12Met), rs766209304, ClinGen CA8643645, cosmic curated COSV10876, ClinVar RCV000294427, REVEL 0.32, CADD 2.38, Conflicting interpretations, not provided; Autosomal recessive limb-girdle muscular dystrophy type 2D
- V12V (p.Val12Val), rs998483886, gnomAD 17-50166076-G-C, CADD 3.63
- V13D (p.Val13Asp), TOPMed rs1354641049, gnomAD rs1354641049, REVEL 0.54, CADD 16.60
- V13I (p.Val13Ile), rs2509114033, ClinGen CA400210778, ClinVar RCV002281541, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- L14F (p.Leu14Phe), Ensembl rs1904980546, REVEL 0.37, CADD 16.40
- L15V (p.Leu15Val), ExAC rs748856279, TOPMed rs748856279, gnomAD rs748856279, REVEL 0.34, CADD 11.60
- L15del (p.Leu15del), rs1345929320, gnomAD 17-50167369-TCTC-, CADD 14.70
- A16S (p.Ala16Ser), gnomAD 17-50167376-G-T, REVEL 0.36, CADD 15.30
- G17R (p.Gly17Arg), rs573792379, ClinGen CA8643683, cosmic curated COSV56250, ClinVar RCV000648062, REVEL 0.30, CADD 9.38, Conflicting interpretations, not provided; Autosomal recessive limb-girdle muscular dystrophy type 2D
- G17E (p.Gly17Glu), gnomAD 17-50167380-G-A, REVEL 0.47, CADD 12.80
- G17G (p.Gly17Gly), gnomAD 17-50167381-G-T, CADD 1.35
- L18V (p.Leu18Val), rs1555568100, ClinGen CA400176338, ClinVar RCV000539687, Ensembl rs1555568100, AlphaMissense 0.09, MetaLR 0.80, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- G19E (p.Gly19Glu), rs774107033, ClinGen CA8643684, ClinVar RCV002899361, ExAC rs774107033, REVEL 0.43, CADD 16.30, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- G19G (p.Gly19Gly), rs2144493078, gnomAD 17-50167387-G-A, CADD 5.30
- D20N (p.Asp20Asn), rs759284746, ClinGen CA8643685, ClinVar RCV000528429, ClinVar RCV000852721, REVEL 0.20, CADD 9.05, Conflicting interpretations, Inborn genetic diseases; Arrhythmogenic right ventricular cardiomyopathy; Autoso
- D20Y (p.Asp20Tyr), rs759284746, ClinGen CA400176375, ClinVar RCV000729954, ClinVar RCV001855744, REVEL 0.38, CADD 19.60, Uncertain significance, not provided; Autosomal recessive limb-girdle muscular dystrophy type 2D
- D20T (p.Asp20Thr), rs1213781897, gnomAD 17-50167383-TG-T, CADD 23.10
- D20G (p.Asp20Gly), gnomAD 17-50167389-A-G, REVEL 0.16, CADD 0.18
- T21I (p.Thr21Ile), rs199804735, ClinGen CA8643686, ClinVar RCV000252821, ClinVar RCV000726346, REVEL 0.26, CADD 2.95, Conflicting interpretations, Inborn genetic diseases; not provided; not specified
- T21S (p.Thr21Ser), gnomAD rs1195821571
- T21T (p.Thr21Thr), rs775361706, gnomAD 17-50167393-C-T, CADD 0.33
- E22K (p.Glu22Lys), rs753784732, ClinGen CA291535971, cosmic curated COSV56251, ClinVar RCV001241464, REVEL 0.31, CADD 3.76, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- A23D (p.Ala23Asp), rs760528436, ClinGen CA400176450, cosmic curated COSV56249, ClinVar RCV003129232, REVEL 0.71, CADD 20.60, Uncertain significance, not provided
- A23G (p.Ala23Gly), ExAC rs760528436, gnomAD rs760528436, REVEL 0.39, CADD 15.70, Uncertain significance
- A23V (p.Ala23Val), ExAC rs760528436, gnomAD rs760528436, REVEL 0.48, CADD 19.50, Uncertain significance
- A23T (p.Ala23Thr), gnomAD 17-50167397-G-A, REVEL 0.30, CADD 15.60
- Q24* (p.Gln24Ter), rs2144493135, ClinGen CA400176463, ClinVar RCV001380121, Ensembl rs2144493135, Pathogenic
- Q24R (p.Gln24Arg), rs2509117878, ClinGen CA2576316717, ClinVar RCV003472665, Likely pathogenic
- Q24Q (p.Gln24Gln), rs1904984718, gnomAD 17-50167402-G-A, CADD 10.40
- Q25* (p.Gln25Ter), gnomAD rs1408325793, CADD 34.00
- Q25K (p.Gln25Lys), gnomAD rs1408325793, REVEL 0.41, CADD 11.70
- T27K (p.Thr27Lys), 1000Genomes rs565069721, ExAC rs565069721, TOPMed rs565069721, gnomAD rs565069721, Likely benign
- T27M (p.Thr27Met), rs565069721, ClinGen CA8643689, cosmic curated COSV56248, ClinVar RCV000328161, REVEL 0.41, CADD 20.20, Conflicting interpretations, Sarcoglycanopathy; not provided; Autosomal recessive limb-girdle muscular dystro
- T27T (p.Thr27Thr), rs2144493184, gnomAD 17-50167411-G-A, CADD 3.84
- L28T (p.Leu28Thr), rs1009354113, gnomAD 17-50167411-GCTAC, CADD 23.10
- L28L (p.Leu28Leu), rs753896716, gnomAD 17-50167412-C-T, CADD 8.63
- H29L (p.His29Leu), rs1387802849, ClinGen CA400176566, ClinVar RCV000786065, gnomAD rs1387802849, REVEL 0.36, CADD 13.50, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- H29Y (p.His29Tyr), rs1555568133, ClinGen CA400176558, ClinVar RCV000598273, ClinVar RCV005742075, REVEL 0.27, CADD 0.32, Conflicting interpretations, Inborn genetic diseases; not provided
- H29H (p.His29His), rs757371081, gnomAD 17-50167417-C-T, CADD 4.47
- P30L (p.Pro30Leu), rs886043256, ClinGen CA10605299, ClinVar RCV000383578, ClinVar RCV002521943, REVEL 0.60, CADD 19.80, Uncertain significance, not provided; Autosomal recessive limb-girdle muscular dystrophy type 2D
- P30S (p.Pro30Ser), rs1327595249, ClinGen CA400176582, cosmic curated COSV10456, ClinVar RCV000531212, REVEL 0.42, CADD 19.50, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- P30T (p.Pro30Thr), gnomAD rs1327595249, REVEL 0.51, CADD 18.70, Likely pathogenic, in LGMDR3
- P30P (p.Pro30Pro), rs754840688, gnomAD 17-50167420-A-G, CADD 2.66
- L31P (p.Leu31Pro), rs903823830, ClinGen CA291535993, ClinVar RCV000665054, UniProt VAR 010403, REVEL 0.59, CADD 19.40, Pathogenic, Autosomal recessive limb-girdle muscular dystrophy
- V32A (p.Val32Ala), rs1017592342, ClinGen CA291535997, cosmic curated COSV10608, ClinVar RCV001963134, REVEL 0.67, CADD 23.50, Pathogenic/Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- V32L (p.Val32Leu), gnomAD 17-50167424-G-T, REVEL 0.69, CADD 24.50
- V32V (p.Val32Val), gnomAD 17-50167426-G-A, CADD 14.50
- G33R (p.Gly33Arg), gnomAD rs1280326054, REVEL 0.92, CADD 26.30
- G33G (p.Gly33Gly), rs750582302, gnomAD 17-50167429-C-T, CADD 6.43
- R34C (p.Arg34Cys), rs758647756, ClinGen CA210084, NCI-TCGA Cosmic COSV1000, cosmic curated COSV10000, REVEL 0.81, AlphaMissense 0.35, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy
- R34H (p.Arg34His), rs371675217, ClinGen CA199071, NCI-TCGA Cosmic COSV5624, cosmic curated COSV56249, REVEL 0.71, CADD 22.90, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy
- R34L (p.Arg34Leu), rs371675217, NCI-TCGA Cosmic COSV5624, cosmic curated COSV56249, 1000Genomes rs371675217, REVEL 0.64, CADD 19.80, Pathogenic, in LGMDR3
- R34P (p.Arg34Pro), NCI-TCGA Cosmic COSV5624, Variant assessed as somatic; moderate impact., in LGMDR3
- R34S (p.Arg34Ser), rs758647756, ClinGen CA400176636, NCI-TCGA Cosmic COSV1000, ClinVar RCV002019675, AlphaMissense 0.35, MetaLR 0.94, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- V35I (p.Val35Ile), rs140629621, ClinGen CA8643694, ClinVar RCV002910008, ESP rs140629621, REVEL 0.21, CADD 3.29, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- V35V (p.Val35Val), rs1216131418, gnomAD 17-50167435-C-T, CADD 7.41
- F36V (p.Phe36Val), rs1904989565, ClinGen CA400176672, ClinVar RCV001305064, Ensembl rs1904989565, AlphaMissense 0.76, MetaLR 0.97, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- F36Y (p.Phe36Tyr), gnomAD 17-50167437-T-A, REVEL 0.78, CADD 26.10
- F36F (p.Phe36Phe), rs755416307, gnomAD 17-50167438-T-C, CADD 10.30
- V37M (p.Val37Met), gnomAD 17-50167439-G-A, REVEL 0.65, CADD 26.20
- V37L (p.Val37Leu), gnomAD 17-50167439-G-T, REVEL 0.55, CADD 22.60
- V37V (p.Val37Val), rs1567738869, gnomAD 17-50167441-G-A, CADD 8.91
- H38R (p.His38Arg), rs2144493345, ClinGen CA400176722, ClinVar RCV001814459, Ensembl rs2144493345, AlphaMissense 0.22, MetaLR 0.91, Likely pathogenic, Abnormality of the musculature
- H38H (p.His38His), rs1451369268, gnomAD 17-50167444-C-T, CADD 8.50
- T39A (p.Thr39Ala), rs540292629, ClinGen CA8643696, ClinVar RCV001000875, ClinVar RCV002549144, REVEL 0.35, CADD 16.80, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D; Inborn genetic disea
- T39I (p.Thr39Ile), TOPMed rs967710629
- T39N (p.Thr39Asn), gnomAD 17-50167446-C-A, REVEL 0.38, CADD 16.80
- L40W (p.Leu40Trp), gnomAD rs1233096399, REVEL 0.88, CADD 26.00
- D41N (p.Asp41Asn), 1000Genomes rs748694967, ExAC rs748694967, gnomAD rs748694967, REVEL 0.45, CADD 22.70
- H42Y (p.His42Tyr), Ensembl rs1332960166
- H42H (p.His42His), rs1904991745, gnomAD 17-50167456-T-C, CADD 0.38
- H42Q (p.His42Gln), gnomAD 17-50167456-T-G, REVEL 0.22, CADD 0.02
- E43K (p.Glu43Lys), NCI-TCGA Cosmic COSV5624, cosmic curated COSV56249, Variant assessed as somatic; moderate impact.
- E43* (p.Glu43Ter), gnomAD 17-50167457-G-T, CADD 34.00
- T44M (p.Thr44Met), rs770516658, ClinGen CA8643698, ClinVar RCV001340209, ExAC rs770516658, REVEL 0.35, CADD 7.45, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- T44S (p.Thr44Ser), gnomAD 17-50167460-A-T, REVEL 0.31, CADD 0.09
- T44T (p.Thr44Thr), rs886044035, gnomAD 17-50167462-G-A, CADD 5.03
- S47N (p.Ser47Asn), NCI-TCGA Cosmic COSV5624, cosmic curated COSV56249, Variant assessed as somatic; moderate impact.
- S47S (p.Ser47Ser), rs1336059898, gnomAD 17-50167471-C-T, CADD 2.15
- L48F (p.Leu48Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L48L (p.Leu48Leu), gnomAD 17-50167474-T-C, CADD 2.14
- P49S (p.Pro49Ser), gnomAD rs1461861588, REVEL 0.30, CADD 18.60
- P49P (p.Pro49Pro), rs745447270, gnomAD 17-50167477-T-C, CADD 1.70
- E50D (p.Glu50Asp), TOPMed rs1904993356
- E50G (p.Glu50Gly), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- E50K (p.Glu50Lys), Ensembl rs1904993106
- H51L (p.His51Leu), TOPMed rs1444419358, gnomAD rs1444419358, REVEL 0.29, CADD 15.30
- H51N (p.His51Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H51Q (p.His51Gln), gnomAD rs1388555738, REVEL 0.35, CADD 0.44
- H51Y (p.His51Tyr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H51H (p.His51His), gnomAD 17-50167483-T-C, CADD 0.88
- V52G (p.Val52Gly), rs148132791, ClinGen CA8643701, ClinVar RCV000274468, ClinVar RCV000693652, REVEL 0.26, CADD 5.64, Uncertain significance, not provided; Autosomal recessive limb-girdle muscular dystrophy type 2D
- V52I (p.Val52Ile), TOPMed rs1372589273, REVEL 0.24, CADD 0.36
- V52V (p.Val52Val), gnomAD 17-50167486-C-A, CADD 1.57
- A53S (p.Ala53Ser), rs60407644, ClinGen CA400177022, ClinVar RCV003136639, AlphaMissense 0.07, MetaLR 0.80, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- A53T (p.Ala53Thr), rs60407644, ClinGen CA8643703, cosmic curated COSV56248, ClinVar RCV000298182, REVEL 0.62, AlphaMissense 0.07, Conflicting interpretations, Autosomal recessive limb-girdle muscular dystrophy; not provided; Autosomal rece
- A53G (p.Ala53Gly), gnomAD 17-50167582-C-G, REVEL 0.26, CADD 14.20
- V54I (p.Val54Ile), rs1485826147, ClinGen CA400177124, ClinVar RCV001579255, gnomAD rs1485826147, REVEL 0.14, CADD 10.60, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- V54V (p.Val54Val), rs1905015392, gnomAD 17-50167586-C-T, CADD 5.38
- P55L (p.Pro55Leu), rs1253463418, ClinGen CA400177153, ClinVar RCV002885703, TOPMed rs1253463418, REVEL 0.17, CADD 14.20, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- P55T (p.Pro55Thr), rs759624003, gnomAD 17-50167585-TCC-T, CADD 22.20
- P55P (p.Pro55Pro), gnomAD 17-50167589-A-G, CADD 4.41
- P56L (p.Pro56Leu), ExAC rs761732772, gnomAD rs761732772, REVEL 0.28, CADD 8.93
- P56P (p.Pro56Pro), rs1193836259, gnomAD 17-50167592-C-T, CADD 3.18
- A57S (p.Ala57Ser), ExAC rs769778891, gnomAD rs769778891, Uncertain significance
- A57T (p.Ala57Thr), rs769778891, ClinGen CA8643727, NCI-TCGA Cosmic COSV5625, cosmic curated COSV56251, REVEL 0.16, CADD 0.37, Uncertain significance, not provided; Autosomal recessive limb-girdle muscular dystrophy type 2D
- A57L (p.Ala57Leu), rs1555568264, gnomAD 17-50167589-AC-A, CADD 15.40
- V58I (p.Val58Ile), 1000Genomes rs141953249, ESP rs141953249, ExAC rs141953249, TOPMed rs141953249, REVEL 0.23, CADD 2.85, Uncertain significance
- V58L (p.Val58Leu), rs141953249, ClinGen CA8643728, ClinVar RCV000593466, ClinVar RCV001245320, REVEL 0.18, CADD 3.66, Uncertain significance, Inborn genetic diseases; not provided; Autosomal recessive limb-girdle muscular
- V58V (p.Val58Val), rs1167800537, gnomAD 17-50167598-C-G, CADD 2.45
- H59R (p.His59Arg), Ensembl rs2144494026
- H59Y (p.His59Tyr), gnomAD rs1376279247
- H59Q (p.His59Gln), gnomAD 17-50167601-C-G, REVEL 0.19, CADD 2.86
- H59H (p.His59His), rs199902950, gnomAD 17-50167601-C-T, CADD 1.45
- I60L (p.Ile60Leu), TOPMed rs1446631821, gnomAD rs1446631821, REVEL 0.32, CADD 6.85
- I60V (p.Ile60Val), gnomAD 17-50167602-A-G, REVEL 0.28, CADD 0.17
- I60I (p.Ile60Ile), gnomAD 17-50167604-C-T, CADD 9.47
- T61I (p.Thr61Ile), TOPMed rs1905020608, REVEL 0.75, CADD 22.80, Uncertain significance, Inborn genetic diseases
- Y62* (p.Tyr62Ter), rs766400853, ClinGen CA400177235, ClinVar RCV003334456, ClinGen CA8643729, CADD 34.00, Pathogenic, in LGMDR3
- Y62H (p.Tyr62His), rs2144494074, ClinGen CA400177224, ClinVar RCV001814397, UniProt VAR 010406, AlphaMissense 0.83, MetaLR 0.95, Likely pathogenic, Abnormality of the musculature
- Y62C (p.Tyr62Cys), gnomAD 17-50167609-A-G, REVEL 0.87, CADD 25.80
- H63N (p.His63Asn), Ensembl rs1905021704, Uncertain significance
- H63Y (p.His63Tyr), rs1905021704, ClinGen CA400177243, ClinVar RCV001361257, Ensembl rs1905021704, AlphaMissense 0.21, MetaLR 0.91, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- H63H (p.His63His), rs373770886, gnomAD 17-50167613-C-T, CADD 0.35
- A64T (p.Ala64Thr), rs759692350, ClinGen CA8643731, ClinVar RCV000274092, ClinVar RCV001859727, REVEL 0.55, CADD 23.30, Conflicting interpretations, not provided; Autosomal recessive limb-girdle muscular dystrophy type 2D
- H65P (p.His65Pro), rs2509118693, ClinGen CA400177291, ClinVar RCV003486338, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- H65Q (p.His65Gln), TOPMed rs1905022570
- L66H (p.Leu66His), rs767928766, ClinGen CA501057, ClinVar RCV000384383, ClinVar RCV003137892, REVEL 0.89, CADD 27.10, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy
- L66P (p.Leu66Pro), ExAC rs767928766, TOPMed rs767928766, gnomAD rs767928766, REVEL 0.91, CADD 28.90, Pathogenic
- Q67E (p.Gln67Glu), rs753180048, ClinGen CA8643732, ClinVar RCV001875342, ExAC rs753180048, REVEL 0.43, CADD 21.60, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- Q67* (p.Gln67Ter), gnomAD 17-50167623-C-T, CADD 38.00
- Q67Q (p.Gln67Gln), rs756679424, gnomAD 17-50167625-G-A, CADD 12.00
- G68E (p.Gly68Glu), rs2144494148, ClinGen CA400177350, NCI-TCGA Cosmic COSV5624, cosmic curated COSV56248, AlphaMissense 0.26, MetaLR 0.94, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy
- G68R (p.Gly68Arg), NCI-TCGA Cosmic COSV5624, cosmic curated COSV56248, REVEL 0.81, CADD 28.30, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- H69Y (p.His69Tyr), gnomAD 17-50167629-C-T, REVEL 0.29, CADD 18.20
- H69H (p.His69His), rs778476146, gnomAD 17-50167631-C-T, CADD 12.00
- P70R (p.Pro70Arg), rs1555568318, ClinGen CA400177397, ClinVar RCV000499843, Ensembl rs1555568318, REVEL 0.97, CADD 27.80, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- P70S (p.Pro70Ser), rs1348067599, ClinGen CA400177393, ClinVar RCV001884413, gnomAD rs1348067599, REVEL 0.95, CADD 27.10, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- P70L (p.Pro70Leu), gnomAD 17-50167633-C-T, REVEL 0.95, CADD 29.20
- D71V (p.Asp71Val), rs2509118747, ClinGen CA400177411, ClinVar RCV003486341, Uncertain significance, Autosomal recessive limb-girdle muscular dystrophy type 2D
- D71A (p.Asp71Ala), gnomAD 17-50167627-GACAC, CADD 32.00
- D71E (p.Asp71Glu), gnomAD 17-50167637-C-A, REVEL 0.83, CADD 25.20
- L72M (p.Leu72Met), gnomAD rs1234995642, REVEL 0.70, CADD 25.80
- L72L (p.Leu72Leu), rs749873696, gnomAD 17-50167640-G-T, CADD 12.90
- P73L (p.Pro73Leu), TOPMed rs1482631076, gnomAD rs1482631076, REVEL 0.96, AlphaMissense 0.70, Conflicting interpretations, not specified; Autosomal recessive limb-girdle muscular dystrophy type 2D
- P73R (p.Pro73Arg), rs1482631076, ClinGen CA400177449, ClinVar RCV002727063, AlphaMissense 0.70, MetaLR 0.99, Pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- P73S (p.Pro73Ser), rs2509118765, ClinGen CA400177443, ClinVar RCV003623429, REVEL 0.93, CADD 26.80, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- P73P (p.Pro73Pro), gnomAD 17-50167643-C-T, CADD 7.80
- R74P (p.Arg74Pro), rs779439298, ClinGen CA400177466, ClinVar RCV002002976, ExAC rs779439298, REVEL 0.73, CADD 24.00, Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy type 2D
- R74Q (p.Arg74Gln), rs779439298, ClinGen CA8643736, NCI-TCGA Cosmic COSV5624, cosmic curated COSV56249, REVEL 0.38, CADD 22.10, Conflicting interpretations, Autosomal recessive limb-girdle muscular dystrophy type 2D
- R74W (p.Arg74Trp), rs757888349, ClinGen CA199069, ClinVar RCV000169146, ClinVar RCV003330528, REVEL 0.75, CADD 24.40, Pathogenic/Likely pathogenic, Autosomal recessive limb-girdle muscular dystrophy; Autosomal recessive limb-gir
- R74L (p.Arg74Leu), gnomAD 17-50167644-C-CTA, CADD 25.00
- p.Arg74delinsLeuThrHisPheSerAspV, gnomAD 17-50167644-C-CTA, CADD 24.90
- R74R (p.Arg74Arg), gnomAD 17-50167646-G-A, CADD 10.60
- W75C (p.Trp75Cys), rs2509118810, ClinGen CA2580094135, ClinVar RCV002880920, Pathogenic
- W75S (p.Trp75Ser), gnomAD 17-50167648-G-C, REVEL 0.98, CADD 32.00
- W75* (p.Trp75Ter), gnomAD 17-50167649-G-A, CADD 39.00
Public SGCA analysis runs
- SGCA analysis run — SGCA (684 variants) — completed 2026-08-21