SELENON (Selenoprotein N) variants and mutations
SELENON (also known as Selenoprotein N) is a human protein-coding gene encoding a selenoprotein N protein. It helps maintain redox and calcium homeostasis within the endoplasmic reticulum of skeletal muscle, particularly during oxidative and mechanical stress. Biallelic loss-of-function variants cause SELENON-related myopathy, often with axial weakness, rigid spine, and disproportionate respiratory impairment. This analysis covers 28 SELENON variants and mutations. Of these, 96% have computational variant effect predictions. Disease context includes rigid spine muscular dystrophy 1, classic multiminicore myopathy, and congenital fiber-type disproportion myopathy. Example SELENON variants include G2C, G2S, and G2V.
Variant analysis overview
- Gene: SELENON
- Protein: Selenoprotein N
- UniProt accession: Q9NZV5
- Organism: Homo sapiens
- Variants analyzed: 28
- Variant scope: all variants
- Completed: 2026-08-22
Variant and mutation evidence
- Variant composition: 13 unspecified-consequence records; 3 frameshift variants; 9 missense variants; 2 synonymous variants; 1 substitution
- Prediction scores: 27 variants have prediction scores (96% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: rigid spine muscular dystrophy 1, classic multiminicore myopathy, congenital fiber-type disproportion myopathy, SELENON-related myopathy, Joubert syndrome and related disorders, hereditary disease, muscular dystrophy, myopathy, rigid spine syndrome, desmin-related myopathy with Mallory body-like inclusions, cleft lip/palate, Abnormality of the musculature.
Protein structure and variant hotspots
- Protein features: 1 domains; 5 post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable SELENON variants
Examples include G2C, G2S, G2V, G2D, G2A, G2G, R3R, R3W. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- G2C (p.Gly2Cys), rs982364753, gnomAD 1-25800234-G-T, REVEL 0.30, MetaLR 0.47
- G2S (p.Gly2Ser), gnomAD 1-25800234-G-A, REVEL 0.26, MetaLR 0.36
- G2V (p.Gly2Val), gnomAD 1-25800235-G-T, REVEL 0.24, MetaLR 0.35
- G2D (p.Gly2Asp), rs1435172502, gnomAD 1-25800235-G-A, REVEL 0.28, MetaLR 0.40
- G2A (p.Gly2Ala), gnomAD 1-25800235-G-C, REVEL 0.22, MetaLR 0.34
- G2G (p.Gly2Gly), rs2047847673, gnomAD 1-25800236-C-G, CADD 10.70
- R3R (p.Arg3Arg), rs866566089, gnomAD 1-25800237-C-A, CADD 11.20
- R3W (p.Arg3Trp), rs866566089, gnomAD 1-25800237-C-T, REVEL 0.26, MetaLR 0.37
- R3L (p.Arg3Leu), gnomAD 1-25800238-G-T, REVEL 0.19, MetaLR 0.34
- R3Q (p.Arg3Gln), rs1234911798, gnomAD 1-25800238-G-A, REVEL 0.22, MetaLR 0.29
- R3P (p.Arg3Pro), rs1234911798, gnomAD 1-25800238-G-C, REVEL 0.30, MetaLR 0.37
- R5N (p.Arg5Asn), rs797044621, gnomAD 1-25800233-GGGCCG, CADD 21.50
- Q8P (p.Gln8Pro), rs797044621, gnomAD 1-25800233-G-GGGC, CADD 19.60
- S13G (p.Ser13Gly), rs2047847645, gnomAD 1-25800234-G-GGCC, CADD 19.50
- T137A (p.Thr137Ala), rs35019869, UniProt VAR 038845, REVEL 0.04, MetaLR 0.02, Benign, SEPN1-related disorder; not specified; not provided
- C142Y (p.Cys142Tyr), rs7349185, UniProt VAR 038846, REVEL 0.04, MetaLR 0.00, Benign, SEPN1-related disorder; not specified; not provided
- G273E (p.Gly273Glu), rs121908182, UniProt VAR 019635, AlphaMissense 0.91, MetaLR 0.93, Pathogenic, Eichsfeld type congenital muscular dystrophy
- H293R (p.His293Arg), rs776738184, UniProt VAR 019636, REVEL 0.95, MetaLR 0.88, Pathogenic/Likely pathogenic, SEPN1-related disorder; Eichsfeld type congenital muscular dystrophy
- G315S (p.Gly315Ser), rs121908188, UniProt VAR 019637, REVEL 0.95, MetaLR 0.92, Likely pathogenic, Eichsfeld type congenital muscular dystrophy; Congenital myopathy 4A, autosomal
- N340I (p.Asn340Ile), rs749911126, UniProt VAR 019638, AlphaMissense 0.48, MetaLR 0.88, Pathogenic, in CMYO3
- Q364X, rs886041584, Pathogenic
- W453S (p.Trp453Ser), rs121908186, UniProt VAR 019639, REVEL 0.94, MetaLR 0.89, Likely pathogenic, Eichsfeld type congenital muscular dystrophy
- U462G, rs121908187, UniProt VAR 019640, SIFT 0.54, Pathogenic, in CMYO3
- G463V (p.Gly463Val), UniProt VAR 058462, MetaLR 0.78, MetaSVM 0.71, Pathogenic, in CMYO3
- R466Q (p.Arg466Gln), rs121908185, UniProt VAR 019641, REVEL 0.73, MetaLR 0.63, Pathogenic/Likely pathogenic, SEPN1-related disorder; Muscular dystrophy; Inborn genetic diseases
- R469Q (p.Arg469Gln), rs779162837, UniProt VAR 058463, REVEL 0.87, MetaLR 0.75, Pathogenic/Likely pathogenic, not provided; Eichsfeld type congenital muscular dystrophy
- R469W (p.Arg469Trp), rs756927098, UniProt VAR 058464, REVEL 0.93, MetaLR 0.86, Pathogenic/Likely pathogenic, not provided; Eichsfeld type congenital muscular dystrophy
- N502K (p.Asn502Lys), rs2294228, UniProt VAR 038847, REVEL 0.09, MetaLR 0.00, Benign, SEPN1-related disorder; not specified; not provided
Public SELENON analysis runs
- SELENON analysis run — SELENON (28 variants) — completed 2026-08-22