SDHD (O14521) variants and mutations
SDHD (also known as O14521) is a human protein-coding gene encoding a succinate dehydrogenase [ubiquinone] cytochrome b small subunit, mitochondrial protein. It provides a membrane-anchoring component of succinate dehydrogenase and is required for normal complex II electron transfer. Germline loss-of-function variants, often showing a parent-of-origin effect, strongly predispose to head-and-neck paragangliomas and pheochromocytomas. This analysis covers 517 SDHD variants and mutations. Of these, 79% have computational variant effect predictions. Disease context includes pheochromocytoma/paraganglioma syndrome 1, hereditary pheochromocytoma-paraganglioma, and paragangliomas with sensorineural hearing loss. Example SDHD variants include M1I, M1L, and M1T.
Variant analysis overview
- Gene: SDHD
- Protein: O14521
- UniProt accession: O14521
- Organism: Homo sapiens
- Variants analyzed: 517
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 440 unspecified-consequence records; 37 synonymous variants; 9 frameshift variants; 23 missense variants; 4 splice-region variants; 3 in-frame deletions; 1 in-frame insertions; 5 substitution
- Prediction scores: 409 variants have prediction scores (79% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: pheochromocytoma/paraganglioma syndrome 1, hereditary pheochromocytoma-paraganglioma, paragangliomas with sensorineural hearing loss, Carney-Stratakis syndrome, pheochromocytoma, mitochondrial complex 2 deficiency, nuclear type 3, Cowden syndrome 3, mitochondrial complex II deficiency, nuclear type 1, Cowden disease, Inherited cancer-predisposing syndrome, hereditary neoplastic syndrome, carcinoid tumor.
Protein structure and variant hotspots
- Protein features: 3 transmembrane segments; 2 binding sites.
- Structural context: 192 variants have structural context.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable SDHD variants
Examples include M1I, M1L, M1T, M1V, A2E, A2G, A2T, A2V. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1I (p.Met1Ile), rs80338842, ClinGen CA016987, ClinVar RCV000007315, ClinVar RCV000020522, MetaLR 0.94, MetaSVM 1.06, Pathogenic, Pheochromocytoma; Carney-Stratakis syndrome; Paragangliomas with sensorineural h
- M1L (p.Met1Leu), rs104894307, ClinGen CA070834, ClinVar RCV000485004, ClinVar RCV000492287, MetaLR 0.94, MetaSVM 1.06, Pathogenic, Hereditary cancer-predisposing syndrome; not provided; Pheochromocytoma
- M1T (p.Met1Thr), rs2498895308, ClinGen CA382616601, ClinVar RCV003783589, Pathogenic, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Carney-Stratak
- M1V (p.Met1Val), rs104894307, ClinGen CA016859, ClinVar RCV002228010, ClinVar RCV004018582, MetaLR 0.94, MetaSVM 1.06, Pathogenic, Pheochromocytoma; Cowden syndrome 3; Carney-Stratakis syndrome
- A2E (p.Ala2Glu), rs1440670464, ClinGen CA382616616, ClinVar RCV004012458, AlphaMissense 0.24, MetaLR 0.78, Uncertain significance, Hereditary pheochromocytoma and paraganglioma
- A2G (p.Ala2Gly), rs1440670464, ClinGen CA382616614, ClinVar RCV002533666, gnomAD rs1440670464, AlphaMissense 0.24, MetaLR 0.78, Uncertain significance, Carney-Stratakis syndrome; Pheochromocytoma; Paragangliomas with sensorineural h
- A2T (p.Ala2Thr), rs1401420432, ClinGen CA382616609, ClinVar RCV002534673, gnomAD rs1401420432, REVEL 0.55, CADD 28.70, Uncertain significance, Paragangliomas with sensorineural hearing loss; Cowden syndrome 3; Carney-Strata
- A2V (p.Ala2Val), rs1440670464, ClinGen CA382616615, cosmic curated COSV54778, ClinVar RCV002240475, REVEL 0.49, AlphaMissense 0.24, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Carney-Stratakis syndrome
- V3A (p.Val3Ala), rs1308232344, ClinGen CA382616626, ClinVar RCV004508400, gnomAD rs1308232344, AlphaMissense 0.06, MetaLR 0.72, Uncertain significance, Hereditary cancer-predisposing syndrome
- V3D (p.Val3Asp), gnomAD rs1308232344, Uncertain significance
- V3F (p.Val3Phe), rs1555186656, ClinGen CA382616622, ClinVar RCV002526129, ClinVar RCV005268658, REVEL 0.53, AlphaMissense 0.10, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- V3G (p.Val3Gly), gnomAD rs1308232344, Uncertain significance
- V3I (p.Val3Ile), rs1555186656, ClinGen CA382616618, ClinVar RCV001962239, Ensembl rs1555186656, AlphaMissense 0.10, MetaLR 0.68, Uncertain significance, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Carney-Stratak
- V3L (p.Val3Leu), rs1555186656, ClinGen CA382616620, ClinVar RCV001921465, Ensembl rs1555186656, AlphaMissense 0.10, MetaLR 0.68, Uncertain significance, Paragangliomas with sensorineural hearing loss; Carney-Stratakis syndrome; Cowde
- V3V (p.Val3Val), gnomAD 11-112086916-T-C, CADD 8.06
- L4F (p.Leu4Phe), rs1032016970, ClinGen CA228550342, NCI-TCGA Cosmic COSV5477, cosmic curated COSV54778, REVEL 0.57, AlphaMissense 0.07, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Paragangliomas with sensorineural hearing l
- L4I (p.Leu4Ile), rs1032016970, ClinGen CA382616630, ClinVar RCV003792134, ClinVar RCV005000036, AlphaMissense 0.07, MetaLR 0.80, Uncertain significance, not provided; Pheochromocytoma; Cowden syndrome 3
- L4V (p.Leu4Val), rs1032016970, ClinGen CA382616632, ClinVar RCV002430843, ClinVar RCV005227760, AlphaMissense 0.07, MetaLR 0.80, Conflicting interpretations, Pheochromocytoma; Cowden syndrome 3; Carney-Stratakis syndrome
- L4S (p.Leu4Ser), gnomAD 11-112086916-TC-T, CADD 14.20
- L4P (p.Leu4Pro), gnomAD 11-112086918-T-C, REVEL 0.56, CADD 23.70
- L4R (p.Leu4Arg), gnomAD 11-112086918-T-G, REVEL 0.55, CADD 24.00
- W5* (p.Trp5Ter), rs104894310, ClinGen CA016834, ClinVar RCV001851719, ClinVar RCV004018583, Pathogenic
- W5C (p.Trp5Cys), Ensembl rs2135264652
- W5R (p.Trp5Arg), rs778202647, ClinGen CA382616643, ClinVar RCV002389250, ClinVar RCV002509839, REVEL 0.55, CADD 22.20, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- R6G (p.Arg6Gly), rs11547889, ClinGen CA070757, ClinVar RCV002533530, ExAC rs11547889, AlphaMissense 0.12, MetaLR 0.78, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Pheoc
- R6K (p.Arg6Lys), rs770924084, ClinGen CA070801, ClinVar RCV002407887, ClinVar RCV003097253, REVEL 0.48, CADD 20.40, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- R6S (p.Arg6Ser), rs200895313, ClinGen CA382616664, ClinVar RCV002534431, ClinVar RCV003999764, AlphaMissense 0.31, MetaLR 0.75, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Cowde
- R6R (p.Arg6Arg), rs200895313, gnomAD 11-112086925-G-A, AlphaMissense 0.31, MetaLR 0.75
- L7P (p.Leu7Pro), rs1865619523, ClinGen CA382616669, ClinVar RCV001974679, NCI-TCGA TCGA novel, AlphaMissense 0.13, MetaLR 0.91, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Paragangliomas with sensorineural hearing l
- L7Q (p.Leu7Gln), rs1865619523, ClinGen CA382616671, ClinVar RCV002242207, ClinVar RCV004951561, AlphaMissense 0.13, MetaLR 0.91, Uncertain significance, Hereditary cancer-predisposing syndrome; Cowden syndrome 3; Carney-Stratakis syn
- L7R (p.Leu7Arg), rs1865619523, ClinGen CA382616670, ClinVar RCV002241255, ClinVar RCV006256305, REVEL 0.67, AlphaMissense 0.13, Uncertain significance, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Cowden syndrom
- L7L (p.Leu7Leu), rs1337542194, gnomAD 11-112086926-C-T, CADD 12.80
- S8C (p.Ser8Cys), Ensembl rs1865619629, Uncertain significance
- S8G (p.Ser8Gly), rs1865619629, ClinGen CA382616673, ClinVar RCV002240503, ClinVar RCV004030500, REVEL 0.56, CADD 13.90, Uncertain significance, Paragangliomas with sensorineural hearing loss; Pheochromocytoma; Cowden syndrom
- S8I (p.Ser8Ile), 1000Genomes rs558914063, ExAC rs558914063, gnomAD rs558914063, REVEL 0.50, CADD 23.10, Uncertain significance
- S8N (p.Ser8Asn), rs558914063, ClinGen CA382616675, ClinVar RCV002242662, ClinVar RCV002432047, REVEL 0.41, CADD 18.80, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Paragangliomas with sensorineural hearing l
- S8R (p.Ser8Arg), TOPMed rs11550094, gnomAD rs11550094, REVEL 0.56, CADD 22.80, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- A9G (p.Ala9Gly), rs1592777287, ClinGen CA382616683, ClinVar RCV002233821, Ensembl rs1592777287, AlphaMissense 0.08, MetaLR 0.68, Uncertain significance, Carney-Stratakis syndrome; Pheochromocytoma; Paragangliomas with sensorineural h
- A9P (p.Ala9Pro), ExAC rs772671893, TOPMed rs772671893, gnomAD rs772671893, REVEL 0.48, CADD 24.30, Uncertain significance
- A9S (p.Ala9Ser), rs772671893, ClinGen CA070945, ClinVar RCV002234310, ClinVar RCV004027932, REVEL 0.49, CADD 21.80, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- A9T (p.Ala9Thr), rs772671893, ClinGen CA382616679, ClinVar RCV002235908, ClinVar RCV004028656, REVEL 0.46, CADD 22.80, Uncertain significance, Hereditary cancer-predisposing syndrome; Cowden syndrome 3; Pheochromocytoma
- A9V (p.Ala9Val), rs1592777287, ClinGen CA382616682, ClinVar RCV001897777, ClinVar RCV002255697, AlphaMissense 0.08, MetaLR 0.68, Uncertain significance, Carney-Stratakis syndrome; Cowden syndrome 3; Pheochromocytoma
- A9D (p.Ala9Asp), gnomAD 11-112086933-C-A, REVEL 0.53, CADD 20.50
- A9A (p.Ala9Ala), rs1555186670, gnomAD 11-112086934-C-T, CADD 8.12
- V10I (p.Val10Ile), rs1555186671, ClinGen CA382616687, ClinVar RCV002438373, ClinVar RCV002526126, AlphaMissense 0.09, MetaLR 0.62, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- V10L (p.Val10Leu), rs1555186671, ClinGen CA382616689, ClinVar RCV004508395, ClinVar RCV006564833, AlphaMissense 0.09, MetaLR 0.62, Conflicting interpretations, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Carney-Stratak
- C11* (p.Cys11Ter), rs104894309, ClinGen CA016967, ClinVar RCV000007324, ClinVar RCV000221327, Pathogenic
- C11Y (p.Cys11Tyr), Ensembl rs1865620286, Uncertain significance, Hereditary cancer-predisposing syndrome
- C11C (p.Cys11Cys), rs104894309, gnomAD 11-112086940-C-T, CADD 13.30
- G12D (p.Gly12Asp), rs764384503, ClinGen CA071285, ClinVar RCV002528396, ClinVar RCV003476278, REVEL 0.44, AlphaMissense 0.11, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- G12R (p.Gly12Arg), rs34677591, ClinGen CA382616709, ClinVar RCV003061423, AlphaMissense 0.09, MetaLR 0.40, Uncertain significance, Pheochromocytoma; Carney-Stratakis syndrome; Paragangliomas with sensorineural h
- G12S (p.Gly12Ser), rs34677591, ClinGen CA016980, cosmic curated COSV54777, ClinVar RCV000007299, REVEL 0.57, AlphaMissense 0.09, Conflicting interpretations, Mitochondrial complex 2 deficiency, nuclear type 3; Carney-Stratakis syndrome; P
- G12V (p.Gly12Val), rs764384503, ClinGen CA382616715, ClinVar RCV001960997, ExAC rs764384503, AlphaMissense 0.11, MetaLR 0.78, Uncertain significance, Carney-Stratakis syndrome; Cowden syndrome 3; Pheochromocytoma
- A13D (p.Ala13Asp), ExAC rs750080041, TOPMed rs750080041, gnomAD rs750080041, Uncertain significance
- A13G (p.Ala13Gly), rs750080041, ClinGen CA382616724, ClinVar RCV002239340, ExAC rs750080041, AlphaMissense 0.12, MetaLR 0.75, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Paragangliomas with s
- A13S (p.Ala13Ser), rs940936212, ClinGen CA228550401, ClinVar RCV002233051, ClinVar RCV002358819, REVEL 0.45, AlphaMissense 0.09, Uncertain significance, Pheochromocytoma; Carney-Stratakis syndrome; Paragangliomas with sensorineural h
- A13T (p.Ala13Thr), rs940936212, ClinGen CA382616718, ClinVar RCV002533254, Ensembl rs940936212, AlphaMissense 0.09, MetaLR 0.75, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- A13V (p.Ala13Val), rs750080041, ClinGen CA071344, ClinVar RCV002352137, ClinVar RCV002544905, REVEL 0.54, AlphaMissense 0.12, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Cowde
- A13A (p.Ala13Ala), rs1566690237, gnomAD 11-112086946-C-T, CADD 12.10
- L14L (p.Leu14Leu), rs1060503772, gnomAD 11-112086947-C-T, CADD 11.30
- G15A (p.Gly15Ala), rs1865621392, ClinGen CA382616743, ClinVar RCV002241767, ClinVar RCV002327653, AlphaMissense 0.10, MetaLR 0.74, Uncertain significance, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Cowden syndrom
- G15E (p.Gly15Glu), rs1865621392, ClinGen CA382616741, ClinVar RCV003784692, AlphaMissense 0.10, MetaLR 0.74, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Pheoc
- G15R (p.Gly15Arg), rs1476121898, ClinGen CA382616736, ClinVar RCV002235295, gnomAD rs1476121898, REVEL 0.51, AlphaMissense 0.10, Uncertain significance, Hereditary cancer-predisposing syndrome; Carney-Stratakis syndrome; Cowden syndr
- G15V (p.Gly15Val), gnomAD 11-112086951-G-T, REVEL 0.50, CADD 32.00
- G16A (p.Gly16Ala), Ensembl rs2135264810
- G16C (p.Gly16Cys), rs1555186687, ClinGen CA382616751, ClinVar RCV001853704, ClinVar RCV003139772, REVEL 0.61, CADD 23.90, Uncertain significance, not provided; Pheochromocytoma; Carney-Stratakis syndrome
- G16D (p.Gly16Asp), rs2135264810, ClinGen CA382616752, ClinVar RCV003781953, ClinVar RCV004673975, AlphaMissense 0.08, MetaLR 0.70, Uncertain significance, Hereditary cancer-predisposing syndrome; Carney-Stratakis syndrome; Paragangliom
- G16R (p.Gly16Arg), rs1555186687, ClinGen CA382616749, ClinVar RCV002526128, ClinVar RCV004722893, REVEL 0.51, CADD 21.30, Uncertain significance, Pheochromocytoma; Carney-Stratakis syndrome; Cowden syndrome 3
- G16V (p.Gly16Val), rs2135264810, ClinGen CA382616756, ClinVar RCV003802662, ClinVar RCV004950689, AlphaMissense 0.08, MetaLR 0.70, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Carney-Stratakis syndrome
- G16G (p.Gly16Gly), rs1555186688, gnomAD 11-112086955-C-T, CADD 14.30
- R17* (p.Arg17Ter), rs1314133983, ClinGen CA382616759, ClinVar RCV002334687, ClinVar RCV002540717, AlphaMissense 0.08, MetaLR 0.67, Pathogenic
- R17G (p.Arg17Gly), rs1314133983, ClinGen CA382616758, ClinVar RCV001819909, ClinVar RCV002241392, REVEL 0.57, AlphaMissense 0.08, Uncertain significance, Carney-Stratakis syndrome; Pheochromocytoma; Cowden syndrome 3
- R17L (p.Arg17Leu), TOPMed rs1865621723, Uncertain significance, Hereditary cancer-predisposing syndrome
- R17P (p.Arg17Pro), NCI-TCGA Cosmic COSV5477, cosmic curated COSV54778, Variant assessed as somatic; moderate impact.
- R17Q (p.Arg17Gln), rs1865621723, ClinGen CA382616761, ClinVar RCV002242695, TOPMed rs1865621723, REVEL 0.52, CADD 23.20, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Pheoc
- R17R (p.Arg17Arg), rs199890548, gnomAD 11-112086958-A-C, CADD 24.20
- A18T (p.Ala18Thr), Ensembl rs2135264839
- A18V (p.Ala18Val), rs192332761, ClinGen CA071521, cosmic curated COSV99736, ClinVar RCV000344579, REVEL 0.48, CADD 23.50, Uncertain significance, Hereditary cancer-predisposing syndrome; Paragangliomas with sensorineural heari
- A18D (p.Ala18Asp), gnomAD 11-112087857-C-A, REVEL 0.72, CADD 23.70
- L19M (p.Leu19Met), Ensembl rs2135266946
- L19P (p.Leu19Pro), rs574698019, ClinGen CA071527, ClinVar RCV001928163, ClinVar RCV003167166, REVEL 0.56, CADD 23.50, Uncertain significance, Carney-Stratakis syndrome; Cowden syndrome 3; Pheochromocytoma
- L19S (p.Leu19Ser), rs886041237, gnomAD 11-112087856-G-GC, CADD 35.00
- L19V (p.Leu19Val), gnomAD 11-112087859-C-G, REVEL 0.45, CADD 17.70
- L19L (p.Leu19Leu), gnomAD 11-112087859-C-T, CADD 14.70
- L20M (p.Leu20Met), rs1298878168, ClinGen CA382616911, ClinVar RCV002563854, gnomAD rs1298878168, AlphaMissense 0.13, MetaLR 0.62, Uncertain significance, Carney-Stratakis syndrome; Pheochromocytoma; Paragangliomas with sensorineural h
- L20S (p.Leu20Ser), rs1865651130, ClinGen CA382616913, ClinVar RCV002357958, REVEL 0.47, CADD 22.80, Uncertain significance, Hereditary cancer-predisposing syndrome
- L20W (p.Leu20Trp), TOPMed rs1865651130, Uncertain significance, Hereditary cancer-predisposing syndrome
- L20C (p.Leu20Cys), rs587776649, gnomAD 11-112087860-TG-T, CADD 23.50
- L20L (p.Leu20Leu), rs1298878168, gnomAD 11-112087862-T-C, AlphaMissense 0.13, MetaLR 0.62
- L21F (p.Leu21Phe), rs1592778703, ClinGen CA382616920, ClinVar RCV001024998, ClinVar RCV002236269, REVEL 0.46, CADD 21.10, Uncertain significance, not provided; Carney-Stratakis syndrome; Mitochondrial complex 2 deficiency, nuc
- L21P (p.Leu21Pro), rs2498899441, ClinGen CA382616923, ClinVar RCV003027948, Uncertain significance, Paragangliomas with sensorineural hearing loss; Pheochromocytoma; Cowden syndrom
- R22* (p.Arg22Ter), rs104894306, ClinGen CA016739, ClinVar RCV000007312, ClinVar RCV000193132, CADD 36.00, Pathogenic
- R22P (p.Arg22Pro), rs1555186772, ClinGen CA382616926, ClinVar RCV002604828, ClinVar RCV006292220, AlphaMissense 0.08, MetaLR 0.59, Uncertain significance, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Carney-Stratak
- R22Q (p.Arg22Gln), rs1555186772, ClinGen CA382616925, NCI-TCGA Cosmic COSV5477, cosmic curated COSV54777, REVEL 0.50, AlphaMissense 0.08, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Cowden syndrome 3
- R22R (p.Arg22Arg), rs104894306, gnomAD 11-112087868-C-A, CADD 14.80
- T23I (p.Thr23Ile), gnomAD 11-112087872-C-T, REVEL 0.48, CADD 16.40
- P24A (p.Pro24Ala), ExAC rs775986509, gnomAD rs775986509, REVEL 0.53, AlphaMissense 0.06, Uncertain significance, Hereditary cancer-predisposing syndrome
- P24L (p.Pro24Leu), rs1865651909, ClinGen CA382616937, ClinVar RCV001920137, ClinVar RCV005729579, AlphaMissense 0.11, MetaLR 0.55, Uncertain significance, Hereditary cancer-predisposing syndrome; Carney-Stratakis syndrome; Pheochromocy
- P24S (p.Pro24Ser), rs775986509, ClinGen CA382616935, ClinVar RCV002005249, ClinVar RCV002361328, AlphaMissense 0.06, MetaLR 0.60, Conflicting interpretations, Carney-Stratakis syndrome; Cowden syndrome 3; Pheochromocytoma
- P24P (p.Pro24Pro), rs1413100881, gnomAD 11-112087876-A-G, CADD 7.69
- V25L (p.Val25Leu), rs878854597, ClinGen CA10582868, ClinVar RCV002229353, ClinVar RCV002378990, AlphaMissense 0.12, MetaLR 0.64, Uncertain significance, Carney-Stratakis syndrome; Pheochromocytoma; Paragangliomas with sensorineural h
- V25V (p.Val25Val), gnomAD 11-112087879-G-A, CADD 14.20
- V26S (p.Val26Ser), gnomAD 11-112087878-TG-T, CADD 26.10
- V26V (p.Val26Val), gnomAD 11-112087882-C-A, CADD 12.50
- R27K (p.Arg27Lys), rs200671534, ClinGen CA071556, ClinVar RCV000401338, ClinVar RCV000570227, REVEL 0.52, CADD 21.00, Benign/Likely benign, Cowden syndrome 3; Pheochromocytoma; Carney-Stratakis syndrome
- R27T (p.Arg27Thr), NCI-TCGA Cosmic COSV5477, cosmic curated COSV54778, Uncertain significance, Hereditary cancer-predisposing syndrome
- P28A (p.Pro28Ala), rs541477171, ClinGen CA382616957, ClinVar RCV002544660, 1000Genomes rs541477171, AlphaMissense 0.10, MetaLR 0.65, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Carney-Stratakis syndrome
- P28H (p.Pro28His), rs2135267114, ClinGen CA382616958, ClinVar RCV001937267, ClinVar RCV004009216, AlphaMissense 0.19, MetaLR 0.68, Uncertain significance, Carney-Stratakis syndrome; Cowden syndrome 3; Pheochromocytoma
- P28S (p.Pro28Ser), rs541477171, ClinGen CA071562, ClinVar RCV001876289, ClinVar RCV002429890, REVEL 0.58, AlphaMissense 0.10, Uncertain significance, Carney-Stratakis syndrome; Pheochromocytoma; Paragangliomas with sensorineural h
- P28T (p.Pro28Thr), rs541477171, ClinGen CA382616956, ClinVar RCV002231791, ClinVar RCV002431616, REVEL 0.76, AlphaMissense 0.10, Uncertain significance, Hereditary cancer-predisposing syndrome; Mitochondrial complex 2 deficiency, nuc
- P28L (p.Pro28Leu), gnomAD 11-112087887-C-T, REVEL 0.71, CADD 26.20
- A29P (p.Ala29Pro), rs776930864, ClinGen CA071569, ClinVar RCV001775826, ClinVar RCV002230657, REVEL 0.66, CADD 23.60, Uncertain significance, Mitochondrial complex 2 deficiency, nuclear type 3; Hereditary cancer-predisposi
- A29T (p.Ala29Thr), rs776930864, ClinGen CA382616961, ClinVar RCV002715787, ClinVar RCV003167664, REVEL 0.48, CADD 23.30, Uncertain significance, Carney-Stratakis syndrome; Cowden syndrome 3; Pheochromocytoma
- A29V (p.Ala29Val), rs1555186774, ClinGen CA382616965, ClinVar RCV002233495, Ensembl rs1555186774, AlphaMissense 0.09, MetaLR 0.70, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Carney-Stratakis syndrome
- A29A (p.Ala29Ala), gnomAD 11-112087891-T-C, CADD 10.00
- H30N (p.His30Asn), cosmic curated COSV54779, 1000Genomes rs561759202, ExAC rs561759202, TOPMed rs561759202, REVEL 0.38, CADD 9.50, Uncertain significance
- H30P (p.His30Pro), rs1592778803, ClinGen CA16616760, ClinVar RCV002234954, ClinVar RCV002291699, REVEL 0.58, CADD 1.42, Uncertain significance, not provided; Hereditary pheochromocytoma and paraganglioma; Hereditary cancer-p
- H30Y (p.His30Tyr), rs561759202, ClinGen CA071577, cosmic curated COSV54778, ClinVar RCV000575014, REVEL 0.55, CADD 5.50, Uncertain significance, Paragangliomas with sensorineural hearing loss; Pheochromocytoma; Cowden syndrom
- I31M (p.Ile31Met), rs766096986, ClinGen CA382616979, cosmic curated COSV54777, ClinVar RCV002373905, REVEL 0.55, CADD 18.30, Uncertain significance, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Carney-Stratakis synd
- I31V (p.Ile31Val), rs1865653068, ClinGen CA382616974, NCI-TCGA Cosmic COSV5477, cosmic curated COSV54779, REVEL 0.48, CADD 2.12, Conflicting interpretations, Hereditary cancer-predisposing syndrome; Hereditary pheochromocytoma and paragan
- I31L (p.Ile31Leu), gnomAD 11-112087895-A-C, REVEL 0.36, CADD 10.50
- I31T (p.Ile31Thr), gnomAD 11-112087896-T-C, REVEL 0.57, CADD 21.50
- I31I (p.Ile31Ile), rs766096986, gnomAD 11-112087897-C-T, CADD 9.76
- S32* (p.Ser32Ter), rs104894305, ClinGen CA016746, ClinVar RCV000007310, ClinVar RCV000505384, AlphaMissense 0.12, MetaLR 0.62, Pathogenic
- S32A (p.Ser32Ala), rs2498899808, ClinGen CA382616981, ClinVar RCV003806345, Uncertain significance, Cowden syndrome 3; Pheochromocytoma; Paragangliomas with sensorineural hearing l
- S32L (p.Ser32Leu), rs104894305, ClinGen CA382616984, cosmic curated COSV54779, ClinVar RCV001994938, AlphaMissense 0.12, MetaLR 0.62, Uncertain significance, Carney-Stratakis syndrome; Cowden syndrome 3; Pheochromocytoma
- S32S (p.Ser32Ser), gnomAD 11-112087900-A-C, CADD 11.20
- A33E (p.Ala33Glu), rs1566692246, ClinGen CA382616988, ClinVar RCV002806858, AlphaMissense 0.11, MetaLR 0.67, Uncertain significance, Paragangliomas with sensorineural hearing loss; Cowden syndrome 3; Pheochromocyt
- A33T (p.Ala33Thr), rs2135267174, ClinGen CA382616985, ClinVar RCV002030411, Ensembl rs2135267174, AlphaMissense 0.08, MetaLR 0.67, Uncertain significance, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Carney-Stratak
- A33V (p.Ala33Val), rs1566692246, ClinGen CA382616990, ClinVar RCV000760072, Ensembl rs1566692246, AlphaMissense 0.11, MetaLR 0.67, Uncertain significance, not provided
- F34C (p.Phe34Cys), rs141802836, ClinGen CA016754, ClinVar RCV000122008, ClinVar RCV000569765, REVEL 0.69, CADD 24.50, Conflicting interpretations, Paragangliomas with sensorineural hearing loss; Cowden syndrome 3; Pheochromocyt
- F34L (p.Phe34Leu), rs2498899868, ClinGen CA382616996, ClinVar RCV003012168, ClinGen CA382616997, Uncertain significance, Pheochromocytoma; Carney-Stratakis syndrome; Paragangliomas with sensorineural h
- L35P (p.Leu35Pro), rs11547892, ClinGen CA228551096, ClinVar RCV003278395, ClinVar RCV005209609, REVEL 0.64, CADD 24.50, Uncertain significance, Cowden syndrome 3; Carney-Stratakis syndrome; Pheochromocytoma
- Q36* (p.Gln36Ter), rs104894303, ClinGen CA016759, ClinVar RCV000007295, ClinVar RCV000492417, AlphaMissense 0.10, MetaLR 0.66, Pathogenic
- Q36H (p.Gln36His), rs766884646, ClinGen CA070592, ClinVar RCV002241405, ClinVar RCV004010746, REVEL 0.57, CADD 24.00, Uncertain significance, Hereditary cancer-predisposing syndrome; Hereditary pheochromocytoma and paragan
- Q36K (p.Gln36Lys), Ensembl rs104894303, Pathogenic
- Q36P (p.Gln36Pro), rs759143732, ClinGen CA070587, ClinVar RCV002242725, ClinVar RCV002420807, REVEL 0.59, CADD 23.50, Uncertain significance, Hereditary cancer-predisposing syndrome; not provided; Carney-Stratakis syndrome
- Q36R (p.Gln36Arg), rs759143732, ClinGen CA16613211, ClinVar RCV001574655, ClinVar RCV002230193, REVEL 0.63, CADD 24.50, Uncertain significance, Paragangliomas with sensorineural hearing loss; Pheochromocytoma; Cowden syndrom
- D37N (p.Asp37Asn), rs1865654125, ClinGen CA382617008, ClinVar RCV002241941, ClinVar RCV002447331, AlphaMissense 0.09, MetaLR 0.66, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Pheoc
- D37V (p.Asp37Val), rs1865654258, ClinGen CA382617013, ClinVar RCV002240993, ClinVar RCV005480608, AlphaMissense 0.14, MetaLR 0.73, Conflicting interpretations, Paragangliomas with sensorineural hearing loss; Carney-Stratakis syndrome; Cowde
- D37Y (p.Asp37Tyr), rs1865654125, ClinGen CA382617010, ClinVar RCV003177714, AlphaMissense 0.09, MetaLR 0.66, Uncertain significance, Hereditary cancer-predisposing syndrome
- R38* (p.Arg38Ter), rs80338843, ClinGen CA016789, ClinVar RCV000007296, ClinVar RCV000020518, CADD 36.00, Pathogenic
- R38G (p.Arg38Gly), cosmic curated COSV10956, TOPMed rs80338843, gnomAD rs80338843, REVEL 0.53, CADD 22.90, Pathogenic
- R38P (p.Arg38Pro), rs199901239, ClinGen CA228551108, ClinVar RCV002232273, ClinVar RCV003159820, REVEL 0.48, CADD 3.76, Uncertain significance, Paragangliomas with sensorineural hearing loss; Pheochromocytoma; Cowden syndrom
- R38Q (p.Arg38Gln), rs199901239, ClinGen CA382617018, ClinVar RCV002241639, ClinVar RCV002451612, REVEL 0.54, CADD 0.95, Conflicting interpretations, Hereditary cancer-predisposing syndrome; Pheochromocytoma; Paragangliomas with s
- R38R (p.Arg38Arg), rs80338843, gnomAD 11-112087916-C-A, CADD 10.30
- R38L (p.Arg38Leu), gnomAD 11-112087917-G-T, REVEL 0.48, CADD 14.60
- P39H (p.Pro39His), ExAC rs752689382, TOPMed rs752689382, gnomAD rs752689382, Uncertain significance
- P39L (p.Pro39Leu), rs752689382, ClinGen CA382617022, ClinVar RCV001010098, ClinVar RCV001816738, REVEL 0.50, CADD 9.93, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Cowde
- P39R (p.Pro39Arg), ExAC rs752689382, TOPMed rs752689382, gnomAD rs752689382, REVEL 0.56, CADD 9.48, Uncertain significance
- P39S (p.Pro39Ser), rs1043566340, ClinGen CA382617020, ClinVar RCV003798342, AlphaMissense 0.07, MetaLR 0.63, Uncertain significance, Pheochromocytoma; Paragangliomas with sensorineural hearing loss; Carney-Stratak
- P39T (p.Pro39Thr), rs1043566340, ClinGen CA228551109, ClinVar RCV002240510, ClinVar RCV002374967, AlphaMissense 0.07, MetaLR 0.63, Uncertain significance, Paragangliomas with sensorineural hearing loss; Pheochromocytoma; Cowden syndrom
- P39P (p.Pro39Pro), gnomAD 11-112087921-T-A, CADD 6.79
- I40L (p.Ile40Leu), rs146276662, ClinGen CA277884, ClinVar RCV000202919, ClinVar RCV000575031, REVEL 0.50, CADD 0.01, Conflicting interpretations, Mitochondrial complex 2 deficiency, nuclear type 3; Carney-Stratakis syndrome; P
- I40M (p.Ile40Met), rs2135267285, ClinGen CA382617027, ClinVar RCV001886205, Ensembl rs2135267285, AlphaMissense 0.07, MetaLR 0.60, Uncertain significance, Paragangliomas with sensorineural hearing loss; Cowden syndrome 3; Pheochromocyt
- I40T (p.Ile40Thr), rs1592778916, ClinGen CA382617025, ClinVar RCV002535923, ClinVar RCV004027515, REVEL 0.56, CADD 2.70, Conflicting interpretations, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Cowde
- I40V (p.Ile40Val), rs146276662, ClinGen CA070608, ClinVar RCV001584275, ClinVar RCV002232274, REVEL 0.51, CADD 0.01, Uncertain significance, not provided; Hereditary cancer-predisposing syndrome; Pheochromocytoma
- P41A (p.Pro41Ala), rs764006625, ClinGen CA382617028, ClinVar RCV002233052, ClinVar RCV004948515, REVEL 0.58, CADD 14.90, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Carney-Stratakis syndrome
- P41L (p.Pro41Leu), rs753724042, ClinGen CA070627, ClinVar RCV002234755, ClinVar RCV002370133, REVEL 0.62, CADD 17.40, Uncertain significance, not provided; Hereditary cancer-predisposing syndrome; Cowden syndrome 3
- P41S (p.Pro41Ser), rs764006625, ClinGen CA070618, cosmic curated COSV54779, ClinVar RCV002241304, REVEL 0.57, CADD 21.20, Uncertain significance, Pheochromocytoma; Cowden syndrome 3; Paragangliomas with sensorineural hearing l
- P41P (p.Pro41Pro), rs1421985099, gnomAD 11-112087927-A-G, CADD 9.38
- E42* (p.Glu42Ter), rs756995021, ClinGen CA382617034, ClinVar RCV003177713, AlphaMissense 0.09, MetaLR 0.55, Pathogenic
- E42G (p.Glu42Gly), rs2498900089, ClinGen CA382617036, ClinVar RCV003278396, ClinVar RCV003777249, REVEL 0.48, CADD 17.60, Conflicting interpretations, Cowden syndrome 3; Carney-Stratakis syndrome; Pheochromocytoma
- E42K (p.Glu42Lys), rs756995021, ClinGen CA070647, ClinVar RCV001910917, ClinVar RCV002397852, REVEL 0.57, AlphaMissense 0.09, Uncertain significance, Carney-Stratakis syndrome; Pheochromocytoma; Paragangliomas with sensorineural h
- E42Q (p.Glu42Gln), ExAC rs756995021, TOPMed rs756995021, gnomAD rs756995021, Uncertain significance
- W43* (p.Trp43Ter), rs104894308, ClinGen CA016785, ClinVar RCV000007322, ClinVar RCV000222413, Pathogenic
- C44* (p.Cys44Ter), rs2498900134, ClinGen CA382617054, ClinVar RCV003804227, Pathogenic
- C44Y (p.Cys44Tyr), rs1566692479, ClinGen CA382617051, ClinVar RCV002533453, ClinVar RCV003999657, AlphaMissense 0.09, MetaLR 0.71, Uncertain significance, Carney-Stratakis syndrome; Paragangliomas with sensorineural hearing loss; Cowde
- G45E (p.Gly45Glu), NCI-TCGA Cosmic COSV5477, cosmic curated COSV54777, Uncertain significance, Pheochromocytoma; Carney-Stratakis syndrome; Cowden syndrome 3
- G45R (p.Gly45Arg), rs2135267356, ClinGen CA382617056, ClinVar RCV002387681, Ensembl rs2135267356, REVEL 0.50, CADD 23.50, Uncertain significance, Hereditary cancer-predisposing syndrome
- G45V (p.Gly45Val), rs2498900147, ClinGen CA382617059, NCI-TCGA Cosmic COSV5477, ClinVar RCV004014281, Uncertain significance, Hereditary pheochromocytoma and paraganglioma
- V46A (p.Val46Ala), 1000Genomes rs2135267375, REVEL 0.54, AlphaMissense 0.08, Uncertain significance, Hereditary cancer-predisposing syndrome
- V46E (p.Val46Glu), rs2135267375, ClinGen CA382617064, ClinVar RCV002381139, AlphaMissense 0.08, MetaLR 0.56, Uncertain significance, Hereditary cancer-predisposing syndrome
- V46L (p.Val46Leu), rs886047699, ClinGen CA382617063, ClinVar RCV002241862, ClinVar RCV006287384, AlphaMissense 0.10, MetaLR 0.65, Uncertain significance, Hereditary cancer-predisposing syndrome; Carney-Stratakis syndrome; Paragangliom
- V46M (p.Val46Met), rs886047699, ClinGen CA10637220, ClinVar RCV000304784, ClinVar RCV002520673, AlphaMissense 0.10, MetaLR 0.65, Uncertain significance, Cowden syndrome 3; Pheochromocytoma; Carney-Stratakis syndrome
- V46H (p.Val46His), gnomAD 11-112087938-GAGT, CADD 29.90
- V46V (p.Val46Val), rs2135267384, gnomAD 11-112087942-G-A, CADD 2.69
- Q47* (p.Gln47Ter), rs1865655722, ClinGen CA382617069, cosmic curated COSV54778, ClinVar RCV001565798, Pathogenic
- Q47P (p.Gln47Pro), rs899706404, ClinGen CA382617070, ClinVar RCV002389453, AlphaMissense 0.06, MetaLR 0.68, Uncertain significance, Hereditary cancer-predisposing syndrome
- Q47R (p.Gln47Arg), rs899706404, ClinGen CA16605858, ClinVar RCV001011433, ClinVar RCV001813776, REVEL 0.59, AlphaMissense 0.06, Uncertain significance, Hereditary cancer-predisposing syndrome; not provided; not specified
Public SDHD analysis runs
- SDHD analysis run — SDHD (517 variants) — completed 2026-08-21