RPGR (Q92834) variants and mutations
RPGR (also known as Q92834) is a human protein-coding gene encoding a x-linked retinitis pigmentosa GTPase regulator protein. It coordinates protein trafficking through the photoreceptor connecting cilium, which is essential for continual renewal of outer segments. Pathogenic variants are a major cause of X-linked retinitis pigmentosa and can also produce cone-rod dystrophy. This analysis covers 569 RPGR variants and mutations. Of these, 72% have computational variant effect predictions. Disease context includes retinitis pigmentosa, Cone rod dystrophy, and Primary ciliary dyskinesia - retinitis pigmentosa. Example RPGR variants include E3K, E6K, and G12S.
Variant analysis overview
- Gene: RPGR
- Protein: Q92834
- UniProt accession: Q92834
- Organism: Homo sapiens
- Variants analyzed: 569
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 353 unspecified-consequence records; 1 stop retained variant; 38 synonymous variants; 154 missense variants; 4 stop-gained variants; 7 in-frame deletions; 10 frameshift variants; 2 splice-region variants; 1 substitution
- Prediction scores: 408 variants have prediction scores (72% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: retinitis pigmentosa, Cone rod dystrophy, Primary ciliary dyskinesia - retinitis pigmentosa, retinitis pigmentosa 3, RPGR-related retinopathy, primary ciliary dyskinesia, X-linked cone-rod dystrophy 1, Retinal dystrophy, cone-rod dystrophy, X-linked cone-rod dystrophy, retinal disorder, ciliopathy.
Protein structure and variant hotspots
- Protein features: 3 post-translational modification sites.
- PTM context: 2 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable RPGR variants
Examples include E3K, E6K, G12S, A13D, A13V, K29E, D35V, H39R. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- E3K (p.Glu3Lys), cosmic curated COSV10589, CADD 22.70, PolyPhen-2 0.94
- E6K (p.Glu6Lys), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58832, CADD 12.80, PolyPhen-2 0.08, Variant assessed as somatic; moderate impact.
- G12S (p.Gly12Ser), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; moderate impact.
- A13D (p.Ala13Asp), NCI-TCGA Cosmic COSV5883, Variant assessed as somatic; moderate impact.
- A13V (p.Ala13Val), rs1435213397, ClinGen CA412746168, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58839, CADD 25.80, PolyPhen-2 1.00, Uncertain significance, Primary ciliary dyskinesia
- K29E (p.Lys29Glu), cosmic curated COSV10517
- D35V (p.Asp35Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H39R (p.His39Arg), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10013, CADD 0.01, PolyPhen-2 0.02, Variant assessed as somatic; moderate impact.
- L40I (p.Leu40Ile), cosmic curated COSV10014
- L40V (p.Leu40Val), NCI-TCGA Cosmic COSV1001, Variant assessed as somatic; moderate impact.
- S41L (p.Ser41Leu), cosmic curated COSV58836, TOPMed rs2067985937, Likely pathogenic
- C42W (p.Cys42Trp), rs1555968526, ClinGen CA412745785, cosmic curated COSV10882, ClinVar RCV000504753, AlphaMissense 0.97, MetaLR 0.70, Uncertain significance, RPGR-related retinopathy
- G43E (p.Gly43Glu), rs62638630, ClinGen CA226352, ClinVar RCV000085051, ClinVar RCV003534330, AlphaMissense 0.99, MetaLR 0.81, Uncertain significance, RPGR-related retinopathy
- G43R (p.Gly43Arg), rs62638629, ClinGen CA226350, ClinVar RCV000085050, ClinVar RCV006451927, AlphaMissense 0.98, MetaLR 0.81, Uncertain significance, RPGR-related retinopathy
- A48S (p.Ala48Ser), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58836, Variant assessed as somatic; moderate impact.
- V50I (p.Val50Ile), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G52* (p.Gly52Ter), rs281865296, ClinGen CA226368, cosmic curated COSV10014, ClinVar RCV000085062, AlphaMissense 0.11, Pathogenic
- G60V (p.Gly60Val), rs62638634, ClinGen CA226376, ClinVar RCV000010580, ClinVar RCV000085072, AlphaMissense 0.99, MetaLR 1.00, Likely pathogenic, RPGR-related retinopathy
- N62K (p.Asn62Lys), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58832, Variant assessed as somatic; moderate impact.
- W64* (p.Trp64Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- Q66R (p.Gln66Arg), cosmic curated COSV58834, Conflicting interpretations, Retinitis pigmentosa 3; not provided
- L67* (p.Leu67Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- G70E (p.Gly70Glu), cosmic curated COSV10013
- G70R (p.Gly70Arg), cosmic curated COSV58838
- S71L (p.Ser71Leu), cosmic curated COSV10810
- K72Q (p.Lys72Gln), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S73L (p.Ser73Leu), cosmic curated COSV10013
- I75V (p.Ile75Val), rs111631988, ClinGen CA202241, ClinVar RCV000086937, ClinVar RCV000177042, CADD 0.01, PolyPhen-2 0.00, Benign, RPGR-related retinopathy
- S76I (p.Ser76Ile), rs1801685, UniProt VAR 013624
- P78Q (p.Pro78Gln), cosmic curated COSV10014
- P78S (p.Pro78Ser), cosmic curated COSV58837
- A83D (p.Ala83Asp), cosmic curated COSV58835
- P86S (p.Pro86Ser), cosmic curated COSV58833
- K88Q (p.Lys88Gln), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R96M (p.Arg96Met), cosmic curated COSV10014
- H98Q (p.His98Gln), rs62638636, ClinGen CA226404, ClinVar RCV000085094, UniProt VAR 008504, CADD 23.50, PolyPhen-2 0.99, not provided
- T99N (p.Thr99Asn), rs62638637, ClinGen CA412745374, ClinVar RCV003890470, ClinVar RCV005415487, AlphaMissense 0.87, MetaLR 0.87, Pathogenic, Retinitis pigmentosa 3
- T99P (p.Thr99Pro), cosmic curated COSV58839
- S102L (p.Ser102Leu), cosmic curated COSV10014
- T103I (p.Thr103Ile), rs2147285611, ClinGen CA412745351, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58833, AlphaMissense 0.78, MetaLR 0.84, Likely pathogenic, RPGR-related retinopathy
- V108A (p.Val108Ala), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; moderate impact.
- G112D (p.Gly112Asp), rs2067878321, ClinGen CA412745285, cosmic curated COSV58840, ClinVar RCV001073580, AlphaMissense 1.00, MetaLR 1.00, Pathogenic/Likely pathogenic, Primary ciliary dyskinesia; Retinal dystrophy
- G117R (p.Gly117Arg), cosmic curated COSV10589
- G120E (p.Gly120Glu), rs2519895072, ClinGen CA412745228, ClinVar RCV002465099, NCI-TCGA TCGA novel, Uncertain significance, not provided
- G122D (p.Gly122Asp), cosmic curated COSV58835, CADD 23.50, PolyPhen-2 0.92, Pathogenic/Likely pathogenic, Primary ciliary dyskinesia; Retinal dystrophy
- T124I (p.Thr124Ile), rs781213060, NCI-TCGA Cosmic COSV1001, cosmic curated COSV10013, ExAC rs781213060, CADD 18.00, PolyPhen-2 0.57, Variant assessed as somatic; moderate impact.
- E125K (p.Glu125Lys), rs769175863, ClinGen CA10385667, NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, CADD 19.20, PolyPhen-2 0.23, Likely benign, Primary ciliary dyskinesia
- R127G (p.Arg127Gly), rs62638643, ClinGen CA226416, ClinVar RCV000085104, ClinVar RCV001075065, AlphaMissense 0.60, MetaLR 0.64, Conflicting interpretations, Retinal dystrophy; not provided; Primary ciliary dyskinesia
- R127I (p.Arg127Ile), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58834, Variant assessed as somatic; moderate impact., in RP3
- F130C (p.Phe130Cys), rs62638644, ClinGen CA412745161, ClinVar RCV001199761, ClinVar RCV005093039, AlphaMissense 0.82, MetaLR 0.76, Uncertain significance, RPGR-related retinopathy
- H131N (p.His131Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V132I (p.Val132Ile), rs768274240, ClinGen CA10385666, ClinVar RCV001509982, ClinVar RCV003931039, CADD 0.58, PolyPhen-2 0.03, Benign, RPGR-related retinopathy
- S138F (p.Ser138Phe), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; moderate impact.
- Q144H (p.Gln144His), cosmic curated COSV10963
- S146F (p.Ser146Phe), cosmic curated COSV10462
- A147S (p.Ala147Ser), cosmic curated COSV58833
- G148V (p.Gly148Val), cosmic curated COSV58836
- S152L (p.Ser152Leu), UniProt VAR 025949, Pathogenic, in RP3
- A153T (p.Ala153Thr), rs2067875526, ClinGen CA412745012, cosmic curated COSV10014, ClinVar RCV001197969, AlphaMissense 0.54, MetaLR 0.78, Uncertain significance, Retinitis pigmentosa 3
- E157* (p.Glu157Ter), cosmic curated COSV10014
- E157G (p.Glu157Gly), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- E157K (p.Glu157Lys), cosmic curated COSV10810
- G159V (p.Gly159Val), cosmic curated COSV99043
- R160I (p.Arg160Ile), NCI-TCGA Cosmic COSV5883, Variant assessed as somatic; moderate impact.
- R160K (p.Arg160Lys), NCI-TCGA Cosmic COSV5883, Variant assessed as somatic; moderate impact.
- R160T (p.Arg160Thr), cosmic curated COSV58837
- L161H (p.Leu161His), cosmic curated COSV10810
- F162V (p.Phe162Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- M163I (p.Met163Ile), cosmic curated COSV10963
- G165S (p.Gly165Ser), cosmic curated COSV58837
- D166N (p.Asp166Asn), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; moderate impact.
- G173A (p.Gly173Ala), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; moderate impact., in RP3 and RPSRDF
- G173R (p.Gly173Arg), rs137852550, ClinGen CA120805, ClinVar RCV003128227, ClinVar RCV003151715, AlphaMissense 0.98, MetaLR 0.98, Likely pathogenic, RPGR-related retinopathy
- L174* (p.Leu174Ter), cosmic curated COSV10517
- K175T (p.Lys175Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- N176H (p.Asn176His), cosmic curated COSV58837
- N176K (p.Asn176Lys), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- S178T (p.Ser178Thr), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10013, Variant assessed as somatic; moderate impact.
- V182I (p.Val182Ile), cosmic curated COSV58838
- Q184H (p.Gln184His), rs5963403, ClinGen CA10385632, ClinVar RCV000251248, ClinVar RCV000459428, CADD 0.86, PolyPhen-2 0.01, Benign
- K190R (p.Lys190Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V192F (p.Val192Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S193F (p.Ser193Phe), cosmic curated COSV10462
- W194C (p.Trp194Cys), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58833, Variant assessed as somatic; moderate impact.
- W194R (p.Trp194Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G198* (p.Gly198Ter), cosmic curated COSV10014
- G198E (p.Gly198Glu), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10013, NCI-TCGA Cosmic COSV5883, Likely pathogenic, RPGR-related retinopathy
- G198V (p.Gly198Val), NCI-TCGA Cosmic COSV1001, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58832, Variant assessed as somatic; moderate impact.
- A203D (p.Ala203Asp), cosmic curated COSV58833
- G209C (p.Gly209Cys), cosmic curated COSV10014
- G209V (p.Gly209Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- F214S (p.Phe214Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G215V (p.Gly215Val), rs62650218, ClinGen CA226433, ClinVar RCV000085115, ClinVar RCV004815044, AlphaMissense 0.99, MetaLR 1.00, Likely pathogenic, not provided
- K221N (p.Lys221Asn), cosmic curated COSV58835
- K221R (p.Lys221Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G223D (p.Gly223Asp), cosmic curated COSV10810, ExAC rs767436763, gnomAD rs767436763
- L224F (p.Leu224Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G230S (p.Gly230Ser), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58834, CADD 0.01, PolyPhen-2 0.04, Variant assessed as somatic; moderate impact.
- R233K (p.Arg233Lys), cosmic curated COSV10013
- P235S (p.Pro235Ser), rs62638651, ClinGen CA226435, ClinVar RCV000010576, ClinVar RCV000085116, AlphaMissense 0.93, MetaLR 0.99, Uncertain significance, Primary ciliary dyskinesia
- L237P (p.Leu237Pro), NCI-TCGA Cosmic COSV5883, NCI-TCGA Cosmic COSV5884, cosmic curated COSV58840, Variant assessed as somatic; moderate impact.
- L237R (p.Leu237Arg), cosmic curated COSV58838
- P242L (p.Pro242Leu), rs773408909, ClinGen CA10385602, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58833, CADD 18.60, PolyPhen-2 0.07, Uncertain significance, Primary ciliary dyskinesia
- P242T (p.Pro242Thr), cosmic curated COSV58836
- E243D (p.Glu243Asp), cosmic curated COSV10013
- A249V (p.Ala249Val), rs1251721610, ClinGen CA412742584, cosmic curated COSV10014, ClinVar RCV001036209, CADD 23.60, PolyPhen-2 0.77, Uncertain significance, Primary ciliary dyskinesia
- C250R (p.Cys250Arg), rs62650220, ClinGen CA226442, ClinVar RCV000085121, UniProt VAR 008506, AlphaMissense 0.99, MetaLR 0.91, not provided
- C250Y (p.Cys250Tyr), rs1601961064, ClinGen CA412742575, ClinVar RCV000990777, ClinVar RCV002549752, AlphaMissense 0.99, MetaLR 0.89, Pathogenic/Likely pathogenic, not provided; Retinitis pigmentosa; Primary ciliary dyskinesia
- G251D (p.Gly251Asp), rs1555966699, ClinGen CA412742559, ClinVar RCV000536819, ClinVar RCV002464247, AlphaMissense 0.99, MetaLR 0.98, Conflicting interpretations, not provided; Primary ciliary dyskinesia
- V257I (p.Val257Ile), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58839, Variant assessed as somatic; moderate impact.
- L258I (p.Leu258Ile), cosmic curated COSV58832
- T259M (p.Thr259Met), cosmic curated COSV10517, CADD 26.40, PolyPhen-2 0.99
- A262G (p.Ala262Gly), rs138018739, ClinGen CA232823, ClinVar RCV000132612, ClinVar RCV000591311, CADD 6.71, PolyPhen-2 0.04, Benign, RPGR-related retinopathy
- T265A (p.Thr265Ala), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; moderate impact.
- G267E (p.Gly267Glu), UniProt VAR 018063, Likely pathogenic, Primary ciliary dyskinesia
- G267R (p.Gly267Arg), rs2147248035, ClinGen CA412741694, ClinVar RCV001531768, UniProt VAR 026127, AlphaMissense 1.00, MetaLR 1.00, Likely pathogenic, not provided
- G272D (p.Gly272Asp), cosmic curated COSV10736, Likely pathogenic, Primary ciliary dyskinesia
- Q273H (p.Gln273His), rs1390141758, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58832, TOPMed rs1390141758, CADD 22.20, PolyPhen-2 1.00, Variant assessed as somatic; moderate impact.
- L274M (p.Leu274Met), cosmic curated COSV10963
- G275S (p.Gly275Ser), rs62642057, ClinGen CA412741594, ClinVar RCV003030558, ClinVar RCV005638193, AlphaMissense 0.99, MetaLR 0.99, Pathogenic, RPGR-related retinopathy
- L280I (p.Leu280Ile), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; moderate impact.
- E282G (p.Glu282Gly), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58835, Variant assessed as somatic; moderate impact.
- S284* (p.Ser284Ter), cosmic curated COSV58836
- E285* (p.Glu285Ter), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Variant assessed as somatic; high impact., in RP3
- E285G (p.Glu285Gly), UniProt VAR 026128, Pathogenic, in RP3
- P286L (p.Pro286Leu), cosmic curated COSV58841
- I289V (p.Ile289Val), rs62640587, ClinGen CA226452, ClinVar RCV000085129, ClinVar RCV000990776, CADD 0.00, PolyPhen-2 0.02, Benign, RPGR-related retinopathy
- Q295E (p.Gln295Glu), cosmic curated COSV10736
- S298R (p.Ser298Arg), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58832, Variant assessed as somatic; moderate impact.
- S301C (p.Ser301Cys), cosmic curated COSV10810
- S301F (p.Ser301Phe), NCI-TCGA Cosmic COSV5883, Variant assessed as somatic; moderate impact.
- S301Y (p.Ser301Tyr), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58834, Variant assessed as somatic; moderate impact.
- C302R (p.Cys302Arg), rs62640589, ClinGen CA226457, ClinVar RCV000085132, ClinVar RCV001251553, AlphaMissense 0.99, MetaLR 0.92, Likely pathogenic, Retinitis pigmentosa 3
- C302Y (p.Cys302Tyr), rs62640590, ClinGen CA10385580, ClinVar RCV000246205, ClinVar RCV000443150, CADD 23.50, PolyPhen-2 1.00, Conflicting interpretations, Retinal dystrophy; Primary ciliary dyskinesia
- D312N (p.Asp312Asn), UniProt VAR 018065, Uncertain significance, RPGR-related retinopathy
- D312Y (p.Asp312Tyr), UniProt VAR 018066, Uncertain significance, RPGR-related retinopathy
- G314C (p.Gly314Cys), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, NCI-TCGA Cosmic COSV5883, Variant assessed as somatic; moderate impact.
- G314S (p.Gly314Ser), cosmic curated COSV58836, TOPMed rs2067497906, CADD 23.30, PolyPhen-2 1.00
- L315V (p.Leu315Val), cosmic curated COSV10609, TOPMed rs2067497764
- G320R (p.Gly320Arg), rs62640593, ClinGen CA226465, ClinVar RCV000085137, ClinVar RCV004815046, AlphaMissense 0.99, MetaLR 1.00, Uncertain significance, Retinal dystrophy
- R323C (p.Arg323Cys), rs757712647, ClinGen CA327926561, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58833, CADD 28.50, PolyPhen-2 0.99, Uncertain significance, Primary ciliary dyskinesia
- R323H (p.Arg323His), rs2067497181, ClinGen CA412740347, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58833, CADD 25.20, PolyPhen-2 0.98, Uncertain significance, RPGR-related retinopathy
- G325R (p.Gly325Arg), NCI-TCGA TCGA novel, CADD 25.10, PolyPhen-2 1.00, Variant assessed as somatic; moderate impact.
- P340H (p.Pro340His), cosmic curated COSV10014, Uncertain significance, Primary ciliary dyskinesia
- P340S (p.Pro340Ser), cosmic curated COSV58840
- N345D (p.Asn345Asp), rs41305223, ClinGen CA226338, cosmic curated COSV58834, ClinVar RCV000085039, CADD 0.83, PolyPhen-2 0.02, Benign, RPGR-related retinopathy
- N345I (p.Asn345Ile), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10014, Ensembl rs2067496129, Variant assessed as somatic; moderate impact.
- L347* (p.Leu347Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- I350M (p.Ile350Met), cosmic curated COSV58837
- L353F (p.Leu353Phe), NCI-TCGA TCGA novel, CADD 33.00, PolyPhen-2 0.78, Variant assessed as somatic; moderate impact.
- A366D (p.Ala366Asp), cosmic curated COSV58835
- P367S (p.Pro367Ser), rs769641256, ClinGen CA10385543, cosmic curated COSV58832, ClinVar RCV002922088, CADD 23.40, PolyPhen-2 0.83, Uncertain significance, Primary ciliary dyskinesia
- H368D (p.His368Asp), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R369C (p.Arg369Cys), rs768571911, ClinGen CA10385539, NCI-TCGA Cosmic COSV5883, cosmic curated COSV58833, CADD 17.40, PolyPhen-2 0.86, Likely benign, RPGR-related retinopathy
- R369H (p.Arg369His), rs1409862085, ClinGen CA412739996, cosmic curated COSV10881, ClinVar RCV002771162, CADD 0.28, PolyPhen-2 0.07, Likely benign, Primary ciliary dyskinesia
- K373N (p.Lys373Asn), cosmic curated COSV10013
- E374* (p.Glu374Ter), rs62635001, ClinGen CA226344, NCI-TCGA Cosmic COSV1001, cosmic curated COSV10013, AlphaMissense 0.13, MetaLR 0.12, Pathogenic
- F377L (p.Phe377Leu), NCI-TCGA Cosmic COSV5883, CADD 0.09, PolyPhen-2 0.00, Conflicting interpretations, Primary ciliary dyskinesia; not provided
- D378N (p.Asp378Asn), rs866428513, ClinGen CA327925034, cosmic curated COSV58838, ClinVar RCV001942919, CADD 6.09, PolyPhen-2 0.04, Uncertain significance, Primary ciliary dyskinesia
- E379* (p.Glu379Ter), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58832, Variant assessed as somatic; high impact.
- P392L (p.Pro392Leu), rs372004762, ClinGen CA10385526, cosmic curated COSV58832, ClinVar RCV002904911, CADD 14.10, PolyPhen-2 0.02, Conflicting interpretations, Primary ciliary dyskinesia
- Q403* (p.Gln403Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- Q403H (p.Gln403His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R409C (p.Arg409Cys), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58837, TOPMed rs2067448260, gnomAD rs2067448260, CADD 25.20, PolyPhen-2 1.00, Variant assessed as somatic; moderate impact.
- R409H (p.Arg409His), rs746041459, ClinGen CA10385517, cosmic curated COSV58837, ClinVar RCV003053362, CADD 23.30, PolyPhen-2 1.00, Uncertain significance, Primary ciliary dyskinesia
- R409P (p.Arg409Pro), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58836, Variant assessed as somatic; moderate impact.
- R411L (p.Arg411Leu), cosmic curated COSV10013
- R411Q (p.Arg411Gln), rs139594653, NCI-TCGA Cosmic COSV1001, ESP rs139594653, ExAC rs139594653, CADD 23.50, PolyPhen-2 1.00, Uncertain significance, Primary ciliary dyskinesia
- R411W (p.Arg411Trp), rs1267740350, gnomAD rs1267740350, CADD 24.90, PolyPhen-2 1.00, Variant assessed as somatic; moderate impact.
- R412* (p.Arg412Ter), rs1601943268, ClinGen CA412739725, cosmic curated COSV58840, ClinVar RCV000787706, Pathogenic
- R412Q (p.Arg412Gln), rs1044939968, ClinGen CA327924860, NCI-TCGA Cosmic COSV1001, cosmic curated COSV10013, CADD 25.60, PolyPhen-2 0.99, Uncertain significance, Primary ciliary dyskinesia
- R413K (p.Arg413Lys), cosmic curated COSV58834, Uncertain significance, Primary ciliary dyskinesia
- E414* (p.Glu414Ter), cosmic curated COSV58837
- R417M (p.Arg417Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S418F (p.Ser418Phe), NCI-TCGA Cosmic COSV5883, cosmic curated COSV58833, NCI-TCGA Cosmic COSV5884, Variant assessed as somatic; moderate impact.
- S418Y (p.Ser418Tyr), NCI-TCGA Cosmic COSV5883, NCI-TCGA Cosmic COSV5884, cosmic curated COSV58840, Variant assessed as somatic; moderate impact.
- S421P (p.Ser421Pro), NCI-TCGA Cosmic COSV1001, cosmic curated COSV10013, Variant assessed as somatic; moderate impact.
- S421T (p.Ser421Thr), NCI-TCGA Cosmic COSV1001, Variant assessed as somatic; moderate impact.
- M424I (p.Met424Ile), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- M424T (p.Met424Thr), cosmic curated COSV58840, ExAC rs770963251, gnomAD rs770963251, CADD 14.20, PolyPhen-2 0.60
Public RPGR analysis runs
- RPGR analysis run — RPGR (569 variants) — completed 2026-08-21