NPHS1 (Nephrin) variants and mutations
NPHS1 (also known as Nephrin) is a human protein-coding gene encoding a nephrin protein. It forms a key structural and signaling component of the slit diaphragm between glomerular podocyte foot processes. Biallelic loss-of-function variants cause congenital nephrotic syndrome of the Finnish type with massive protein loss beginning early in life. This analysis covers 1,958 NPHS1 variants and mutations. Of these, 77% have computational variant effect predictions. Disease context includes congenital nephrotic syndrome, Finnish type, nephrotic syndrome, and dental enamel hypoplasia. Example NPHS1 variants include M1T, A2T, and A2V.
Variant analysis overview
- Gene: NPHS1
- Protein: Nephrin
- UniProt accession: O60500
- Organism: Homo sapiens
- Variants analyzed: 1958
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 1,729 unspecified-consequence records; 2 in-frame insertions; 90 synonymous variants; 104 missense variants; 18 frameshift variants; 6 stop-gained variants; 3 in-frame deletions; 4 splice-region variants; 2 substitution
- Prediction scores: 1,514 variants have prediction scores (77% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: congenital nephrotic syndrome, Finnish type, nephrotic syndrome, dental enamel hypoplasia, tooth agenesis, focal segmental glomerulosclerosis, familial nephrotic syndrome, hereditary disease, glomerulonephritis, renal dialysis, dental caries, familial idiopathic steroid-resistant nephrotic syndrome, kidney failure.
Protein structure and variant hotspots
- Protein features: 1 transmembrane segments; 9 domains; 15 post-translational modification sites.
- Structural context: 1,255 variants have structural context.
- PTM context: 26 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable NPHS1 variants
Examples include M1T, A2T, A2V, L3M, G4E, G4R, G4V, T5K. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1T (p.Met1Thr), rs942323517, ClinGen CA307791385, ClinVar RCV002681527, MetaLR 0.21, MetaSVM -0.84, Pathogenic/Likely pathogenic, not provided; Finnish congenital nephrotic syndrome
- A2T (p.Ala2Thr), ExAC rs780342009, gnomAD rs780342009, REVEL 0.07, CADD 9.39
- A2V (p.Ala2Val), TOPMed rs1973273450, REVEL 0.11, CADD 17.10
- L3M (p.Leu3Met), rs756995769, ClinGen CA9390949, ClinVar RCV002995252, ExAC rs756995769, REVEL 0.13, CADD 18.60, Likely benign, not provided
- G4E (p.Gly4Glu), 1000Genomes rs557888757, ExAC rs557888757, gnomAD rs557888757, REVEL 0.04, CADD 3.79
- G4R (p.Gly4Arg), rs1338229781, ClinGen CA405412771, ClinVar RCV001578737, gnomAD rs1338229781, AlphaMissense 0.08, MetaLR 0.13, Uncertain significance, Finnish congenital nephrotic syndrome
- G4V (p.Gly4Val), NCI-TCGA TCGA novel, REVEL 0.06, CADD 3.96, Variant assessed as somatic; moderate impact.
- T5K (p.Thr5Lys), 1000Genomes rs191850409, ExAC rs191850409, TOPMed rs191850409, gnomAD rs191850409, REVEL 0.14, CADD 1.16, Likely benign
- T5M (p.Thr5Met), rs191850409, ClinGen CA9390947, cosmic curated COSV10591, ClinVar RCV000907367, REVEL 0.06, CADD 7.48, Conflicting interpretations, Congenital nephrotic syndrome; not provided; Finnish congenital nephrotic syndro
- T5R (p.Thr5Arg), rs2513787438, ClinGen CA2576759101, ClinVar RCV003555126, Pathogenic
- T6K (p.Thr6Lys), 1000Genomes rs150180768, ESP rs150180768, ExAC rs150180768, TOPMed rs150180768, REVEL 0.06, CADD 0.01, Likely benign
- T6M (p.Thr6Met), rs150180768, ClinGen CA9390946, cosmic curated COSV10079, ClinVar RCV003073965, REVEL 0.05, CADD 0.03, Likely benign, Inborn genetic diseases; not provided
- T6R (p.Thr6Arg), rs150180768, ClinGen CA307791360, ClinVar RCV002294639, 1000Genomes rs150180768, REVEL 0.09, CADD 0.01, Uncertain significance, Focal segmental glomerulosclerosis
- L7F (p.Leu7Phe), rs202032966, ClinGen CA405412735, ClinVar RCV002921714, REVEL 0.24, CADD 0.01, Uncertain significance, Inborn genetic diseases
- L7R (p.Leu7Arg), ExAC rs765269906, TOPMed rs765269906, gnomAD rs765269906, REVEL 0.22, CADD 5.70
- L7V (p.Leu7Val), 1000Genomes rs202032966, gnomAD rs202032966, REVEL 0.23, CADD 0.00
- A9D (p.Ala9Asp), TOPMed rs1599848663, gnomAD rs1599848663, REVEL 0.17, CADD 14.00
- A9T (p.Ala9Thr), rs376793744, ClinGen CA9390943, ClinVar RCV000401008, ClinVar RCV001124815, REVEL 0.18, CADD 1.27, Uncertain significance, Inborn genetic diseases; Finnish congenital nephrotic syndrome; not provided
- S10P (p.Ser10Pro), gnomAD rs1476925013, REVEL 0.10, CADD 0.04
- S10Y (p.Ser10Tyr), TOPMed rs914737033
- L12P (p.Leu12Pro), gnomAD rs1200535267, REVEL 0.51, CADD 24.20
- L14P (p.Leu14Pro), rs1060499706, ClinGen CA16609461, ClinVar RCV000449573, Ensembl rs1060499706, REVEL 0.21, CADD 16.70, Uncertain significance, Finnish congenital nephrotic syndrome
- G15E (p.Gly15Glu), rs373782564, ClinGen CA9390941, ClinVar RCV001965555, ClinVar RCV003250350, REVEL 0.15, CADD 11.90, Uncertain significance, not provided; Inborn genetic diseases
- G15R (p.Gly15Arg), rs73928330, ClinGen CA9390942, ClinVar RCV000244392, ClinVar RCV000669644, REVEL 0.13, CADD 16.90, Conflicting interpretations, not specified; not provided; Finnish congenital nephrotic syndrome
- G15V (p.Gly15Val), rs373782564, ESP rs373782564, ExAC rs373782564, TOPMed rs373782564, REVEL 0.12, CADD 11.40, Uncertain significance
- L16V (p.Leu16Val), Ensembl rs1568457956, REVEL 0.20, CADD 8.07
- E19K (p.Glu19Lys), TOPMed rs1973271375, REVEL 0.07, CADD 4.39
- G20D (p.Gly20Asp), TOPMed rs1350656344
- G20S (p.Gly20Ser), TOPMed rs1973271302
- G20V (p.Gly20Val), TOPMed rs1350656344
- L21R (p.Leu21Arg), Ensembl rs1599848322
- A22E (p.Ala22Glu), 1000Genomes rs116617171, ExAC rs116617171, TOPMed rs116617171, gnomAD rs116617171, REVEL 0.20, CADD 18.20, Benign
- A22V (p.Ala22Val), rs116617171, ClinGen CA9390924, cosmic curated COSV62288, ClinVar RCV000490334, REVEL 0.12, CADD 16.50, Conflicting interpretations, not provided; not specified; Finnish congenital nephrotic syndrome
- Q23P (p.Gln23Pro), Ensembl rs1973266553
- L24* (p.Leu24Ter), rs2513786480, ClinGen CA405412453, ClinVar RCV002307169, Likely pathogenic
- L24F (p.Leu24Phe), gnomAD rs1366100934
- A25V (p.Ala25Val), rs368988883, ClinGen CA9390921, cosmic curated COSV10466, ClinVar RCV003562039, REVEL 0.08, CADD 4.76, Likely benign, not provided
- P27L (p.Pro27Leu), Ensembl rs866041948
- A28P (p.Ala28Pro), rs768721706, ClinGen CA9390918, ClinVar RCV002665797, ExAC rs768721706, REVEL 0.17, CADD 16.60, Uncertain significance, Inborn genetic diseases
- A28V (p.Ala28Val), rs2513786392, ClinGen CA405412396, ClinVar RCV003195450, REVEL 0.12, CADD 20.00, Uncertain significance, Inborn genetic diseases
- S29F (p.Ser29Phe), rs1339541913, ClinGen CA405412383, ClinVar RCV001992433, ClinVar RCV002492072, AlphaMissense 0.12, MetaLR 0.36, Uncertain significance, not provided; Finnish congenital nephrotic syndrome
- V30I (p.Val30Ile), cosmic curated COSV62288, ExAC rs770291189, TOPMed rs770291189, gnomAD rs770291189, REVEL 0.05, CADD 1.42
- P31L (p.Pro31Leu), cosmic curated COSV10527, TOPMed rs1015599425, gnomAD rs1015599425, REVEL 0.16, CADD 18.20
- P31S (p.Pro31Ser), TOPMed rs1973265670
- R32Q (p.Arg32Gln), rs781561486, ClinGen CA9390913, cosmic curated COSV62286, ClinVar RCV003990511, REVEL 0.12, CADD 20.50, Uncertain significance, Finnish congenital nephrotic syndrome
- R32W (p.Arg32Trp), rs148104086, ClinGen CA9390914, ClinVar RCV003573358, ESP rs148104086, REVEL 0.47, CADD 25.80, Likely benign, not provided
- G33D (p.Gly33Asp), TOPMed rs1311434081, gnomAD rs1311434081, REVEL 0.08, CADD 16.90
- F34I (p.Phe34Ile), 1000Genomes rs201546612, gnomAD rs201546612, REVEL 0.40, CADD 25.40, Uncertain significance, Finnish congenital nephrotic syndrome
- F34L (p.Phe34Leu), 1000Genomes rs201546612, gnomAD rs201546612, REVEL 0.40, CADD 25.90, Uncertain significance
- F34S (p.Phe34Ser), ExAC rs771678437, gnomAD rs771678437, REVEL 0.62, CADD 27.20
- W35* (p.Trp35Ter), rs1450477596, ClinGen CA405412314, ClinVar RCV001891874, ClinVar RCV003464200, CADD 37.00, Pathogenic
- A36D (p.Ala36Asp), TOPMed rs1973264895
- A36T (p.Ala36Thr), ExAC rs747796960, TOPMed rs747796960, gnomAD rs747796960, REVEL 0.03, CADD 16.10, Uncertain significance, Inborn genetic diseases
- E39K (p.Glu39Lys), rs375670819, ClinGen CA9390910, cosmic curated COSV62287, ClinVar RCV000370301, REVEL 0.05, CADD 20.40, Conflicting interpretations, Focal segmental glomerulosclerosis; Congenital nephrotic syndrome; not provided
- N40S (p.Asn40Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- N40T (p.Asn40Thr), TOPMed rs891201320
- L41P (p.Leu41Pro), gnomAD rs1401704364, REVEL 0.41, CADD 22.70
- T42M (p.Thr42Met), rs754516370, NCI-TCGA Cosmic COSV6228, cosmic curated COSV62287, 1000Genomes rs754516370, REVEL 0.28, CADD 24.70, Uncertain significance, Inborn genetic diseases
- V43A (p.Val43Ala), rs140626538, ClinGen CA9390907, ClinVar RCV000243577, ClinVar RCV000588978, REVEL 0.16, CADD 13.10, Conflicting interpretations, not specified; not provided; Congenital nephrotic syndrome
- V44G (p.Val44Gly), ExAC rs756017240, gnomAD rs756017240, REVEL 0.15, CADD 22.90
- E45D (p.Glu45Asp), ExAC rs757545314, gnomAD rs757545314, REVEL 0.16, CADD 14.90, Likely benign
- E45K (p.Glu45Lys), rs199932050, ClinGen CA9390904, ClinVar RCV003077743, ClinVar RCV004071756, REVEL 0.14, CADD 17.70, Conflicting interpretations, not provided; Inborn genetic diseases
- E45Q (p.Glu45Gln), 1000Genomes rs199932050, ExAC rs199932050, TOPMed rs199932050, gnomAD rs199932050, REVEL 0.09, CADD 16.40, Uncertain significance, Finnish congenital nephrotic syndrome
- G46E (p.Gly46Glu), rs2513786137, ClinGen CA405412184, ClinVar RCV003268492, Uncertain significance, Inborn genetic diseases
- G46R (p.Gly46Arg), TOPMed rs1344500638, REVEL 0.79, CADD 24.60
- A47T (p.Ala47Thr), ExAC rs764249562, TOPMed rs764249562, gnomAD rs764249562, REVEL 0.02, CADD 7.01, Uncertain significance, Finnish congenital nephrotic syndrome
- V49A (p.Val49Ala), TOPMed rs1973263497, gnomAD rs1973263497, REVEL 0.16, CADD 7.69, Uncertain significance
- V49G (p.Val49Gly), rs1973263497, ClinGen CA405412136, ClinVar RCV001810544, TOPMed rs1973263497, REVEL 0.39, CADD 18.70, Uncertain significance, Finnish congenital nephrotic syndrome
- E50A (p.Glu50Ala), TOPMed rs1244719642
- E50D (p.Glu50Asp), ExAC rs760073893, gnomAD rs760073893, REVEL 0.04, CADD 11.70
- E50K (p.Glu50Lys), ExAC rs765675306, gnomAD rs765675306, REVEL 0.04, CADD 9.34
- R52C (p.Arg52Cys), rs1431747804, NCI-TCGA Cosmic COSV1008, cosmic curated COSV10080, gnomAD rs1431747804, REVEL 0.12, CADD 22.80, Variant assessed as somatic; moderate impact.
- R52H (p.Arg52His), rs771076402, ClinGen CA9390894, ClinVar RCV002627824, ExAC rs771076402, REVEL 0.14, CADD 5.34, Likely benign, not provided
- G54E (p.Gly54Glu), ESP rs369112617, TOPMed rs369112617, gnomAD rs369112617, REVEL 0.16, CADD 14.50
- G54R (p.Gly54Arg), ExAC rs774170395, gnomAD rs774170395, REVEL 0.24, CADD 22.70
- G54V (p.Gly54Val), ESP rs369112617, TOPMed rs369112617, gnomAD rs369112617, REVEL 0.22, CADD 22.20
- G54W (p.Gly54Trp), NCI-TCGA Cosmic COSV6228, cosmic curated COSV62289, Variant assessed as somatic; moderate impact.
- V55D (p.Val55Asp), rs2513786002, ClinGen CA2584604473, ClinVar RCV003572094, Pathogenic
- V55F (p.Val55Phe), ExAC rs768382806, TOPMed rs768382806, gnomAD rs768382806
- V55I (p.Val55Ile), ExAC rs768382806, TOPMed rs768382806, gnomAD rs768382806, REVEL 0.19, CADD 23.00
- V55L (p.Val55Leu), ExAC rs768382806, TOPMed rs768382806, gnomAD rs768382806, REVEL 0.24, CADD 23.20
- T57N (p.Thr57Asn), Ensembl rs1599848088, REVEL 0.10, CADD 15.40, Uncertain significance, Finnish congenital nephrotic syndrome
- T57P (p.Thr57Pro), gnomAD rs1441837750, REVEL 0.06, CADD 13.40
- P58L (p.Pro58Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P58R (p.Pro58Arg), TOPMed rs1973262484
- P58S (p.Pro58Ser), cosmic curated COSV62286, TOPMed rs1973262633, REVEL 0.05, CADD 19.60
- G59D (p.Gly59Asp), rs1216664192, NCI-TCGA Cosmic COSV6228, cosmic curated COSV62287, TOPMed rs1216664192, REVEL 0.07, CADD 22.20, Variant assessed as somatic; moderate impact.
- S60G (p.Ser60Gly), Ensembl rs368676192, REVEL 0.09, CADD 16.00
- S60N (p.Ser60Asn), gnomAD rs1167489128, REVEL 0.15, CADD 23.50
- S60R (p.Ser60Arg), Ensembl rs368676192
- A61E (p.Ala61Glu), 1000Genomes rs116620503, ExAC rs116620503, TOPMed rs116620503, gnomAD rs116620503, Likely benign
- A61V (p.Ala61Val), rs116620503, ClinGen CA9390890, cosmic curated COSV62287, ClinVar RCV002127686, REVEL 0.05, CADD 0.23, Likely benign, not provided
- V62A (p.Val62Ala), ExAC rs756068896
- Q63* (p.Gln63Ter), rs2513785885, ClinGen CA405411591, ClinVar RCV002310466, Likely pathogenic
- W64S (p.Trp64Ser), rs386833897, ClinGen CA250153, ClinVar RCV000049868, UniProt VAR 013029, REVEL 0.89, CADD 26.70, Likely pathogenic, Finnish congenital nephrotic syndrome
- A65D (p.Ala65Asp), cosmic curated COSV62287, ExAC rs745815470, gnomAD rs745815470, REVEL 0.26, CADD 25.30
- A65P (p.Ala65Pro), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- A65T (p.Ala65Thr), TOPMed rs1238341218
- D67G (p.Asp67Gly), gnomAD rs1265073873, REVEL 0.20, CADD 27.20
- G68R (p.Gly68Arg), Ensembl rs1472599014
- G68W (p.Gly68Trp), cosmic curated COSV10743, Ensembl rs1472599014
- L70I (p.Leu70Ile), gnomAD rs1487823473, REVEL 0.24, CADD 26.60
- L71P (p.Leu71Pro), rs1568457698, ClinGen CA405411478, ClinVar RCV000712424, Ensembl rs1568457698, AlphaMissense 0.68, MetaLR 0.50, Uncertain significance, not provided
- L71R (p.Leu71Arg), rs2513785791, ClinGen CA2580096903, ClinVar RCV002797368, Pathogenic
- G72C (p.Gly72Cys), Ensembl rs2146832473
- P73L (p.Pro73Leu), rs752777463, ClinGen CA9390881, ClinVar RCV001122044, ClinVar RCV001192700, REVEL 0.41, CADD 28.80, Uncertain significance, not specified; Congenital nephrotic syndrome; not provided
- P73S (p.Pro73Ser), ESP rs376923714, ExAC rs376923714, TOPMed rs376923714, gnomAD rs376923714, REVEL 0.29, CADD 26.40
- D74N (p.Asp74Asn), 1000Genomes rs557710851, ExAC rs557710851, REVEL 0.03, CADD 15.50
- P75L (p.Pro75Leu), cosmic curated COSV10527, TOPMed rs1218451320, gnomAD rs1218451320
- P75S (p.Pro75Ser), TOPMed rs1973260793, REVEL 0.07, CADD 22.50
- P75T (p.Pro75Thr), TOPMed rs1973260793
- R76S (p.Arg76Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R76T (p.Arg76Thr), ExAC rs777175636, gnomAD rs777175636, REVEL 0.02, CADD 15.90
- P78L (p.Pro78Leu), TOPMed rs1295860951, gnomAD rs1295860951, REVEL 0.54, CADD 29.00, Uncertain significance, Finnish congenital nephrotic syndrome
- G79C (p.Gly79Cys), rs2513785693, ClinGen CA405411384, ClinVar RCV002915580, Uncertain significance, Inborn genetic diseases
- G79R (p.Gly79Arg), rs2513785701, ClinGen CA2580096901, ClinVar RCV002307111, Likely pathogenic
- F80L (p.Phe80Leu), Ensembl rs2146832406
- P81L (p.Pro81Leu), ExAC rs761152159, TOPMed rs761152159, gnomAD rs761152159, REVEL 0.24, CADD 24.00
- P81Q (p.Pro81Gln), NCI-TCGA Cosmic COSV1008, cosmic curated COSV10080, REVEL 0.28, CADD 25.30, Variant assessed as somatic; moderate impact.
- P81R (p.Pro81Arg), ExAC rs761152159, TOPMed rs761152159, gnomAD rs761152159, REVEL 0.33, CADD 25.50
- P81S (p.Pro81Ser), gnomAD rs1434933933, REVEL 0.25, CADD 24.10
- Y83* (p.Tyr83Ter), rs386833914, ClinGen CA250190, ClinVar RCV000049888, ClinVar RCV002514255, CADD 29.40, Pathogenic
- Y83C (p.Tyr83Cys), gnomAD rs1425382291, REVEL 0.49, CADD 25.40
- Y83D (p.Tyr83Asp), Ensembl rs1599847925
- R84C (p.Arg84Cys), rs1168071834, ClinGen CA405411344, ClinVar RCV001342337, ClinVar RCV001831084, REVEL 0.32, CADD 25.50, Uncertain significance, not provided
- R84H (p.Arg84His), TOPMed rs959393189, gnomAD rs959393189, REVEL 0.05, CADD 0.15
- R84S (p.Arg84Ser), TOPMed rs1168071834, gnomAD rs1168071834, REVEL 0.07, CADD 15.90, Uncertain significance
- E86A (p.Glu86Ala), TOPMed rs1973259458
- G87E (p.Gly87Glu), ExAC rs748939918, gnomAD rs748939918, REVEL 0.42, CADD 24.80, Uncertain significance, Finnish congenital nephrotic syndrome
- D88E (p.Asp88Glu), rs1973259133, ClinGen CA405411301, ClinVar RCV003728254, Ensembl rs1973259133, REVEL 0.14, CADD 22.40, Uncertain significance, not provided
- D88H (p.Asp88His), gnomAD rs1246225340, REVEL 0.30, CADD 23.40
- D88V (p.Asp88Val), rs1205262136, ClinGen CA405411304, ClinVar RCV002916114, TOPMed rs1205262136, REVEL 0.41, CADD 26.70, Uncertain significance, Inborn genetic diseases
- P89S (p.Pro89Ser), rs1334881131, ClinGen CA405411291, ClinVar RCV004491015, TOPMed rs1334881131, REVEL 0.04, CADD 19.40, Uncertain significance, Inborn genetic diseases
- A90D (p.Ala90Asp), rs1459119408, ClinGen CA405411274, ClinVar RCV004491016, AlphaMissense 0.08, MetaLR 0.21, Uncertain significance, Inborn genetic diseases
- A90G (p.Ala90Gly), gnomAD rs1459119408
- A90S (p.Ala90Ser), TOPMed rs1973258948, REVEL 0.02, CADD 5.43
- A90V (p.Ala90Val), gnomAD rs1459119408, REVEL 0.14, AlphaMissense 0.08
- R91G (p.Arg91Gly), ExAC rs774932492, REVEL 0.11, CADD 21.70
- R91I (p.Arg91Ile), gnomAD rs1256453272, REVEL 0.15, CADD 14.60
- G92=, NCI-TCGA Cosmic COSV1007, Variant assessed as somatic; low impact.
- H95Y (p.His95Tyr), rs761207157, ClinGen CA9390858, ClinVar RCV004491018, ExAC rs761207157, REVEL 0.33, CADD 25.40, Uncertain significance, Inborn genetic diseases
- L96Q (p.Leu96Gln), rs2513785174, ClinGen CA405411125, ClinVar RCV003685149, REVEL 0.86, CADD 30.00, Likely pathogenic, not provided
- L96V (p.Leu96Val), rs386833929, ClinGen CA250214, ClinVar RCV000049903, ClinVar RCV001853056, REVEL 0.71, CADD 26.00, Likely pathogenic, Finnish congenital nephrotic syndrome; not provided
- H97L (p.His97Leu), ExAC rs750879791, TOPMed rs750879791, gnomAD rs750879791, REVEL 0.03, CADD 9.36, Uncertain significance, Inborn genetic diseases
- H97Q (p.His97Gln), ExAC rs767994137, TOPMed rs767994137, gnomAD rs767994137, REVEL 0.04, CADD 1.72, Likely benign
- I98V (p.Ile98Val), Ensembl rs1568457541, REVEL 0.43, CADD 23.90
- E99* (p.Glu99Ter), rs1006352232, ClinGen CA405411075, ClinVar RCV002306992, ClinVar RCV003099160, AlphaMissense 0.08, MetaLR 0.14, Pathogenic
- E99K (p.Glu99Lys), rs1006352232, ClinGen CA307790726, ClinVar RCV003085565, ClinVar RCV003274209, REVEL 0.12, AlphaMissense 0.08, Uncertain significance, Inborn genetic diseases; not provided
- A100S (p.Ala100Ser), rs1379397351, ClinGen CA405411055, ClinVar RCV001122043, TOPMed rs1379397351, AlphaMissense 0.08, MetaLR 0.09, Uncertain significance, Congenital nephrotic syndrome
- A100T (p.Ala100Thr), TOPMed rs1379397351, gnomAD rs1379397351, REVEL 0.07, AlphaMissense 0.08, Uncertain significance
- A100V (p.Ala100Val), Ensembl rs1973253766, REVEL 0.12, CADD 12.00
- C101Y (p.Cys101Tyr), NCI-TCGA Cosmic COSV6228, cosmic curated COSV62288, Variant assessed as somatic; moderate impact.
- D102G (p.Asp102Gly), Ensembl rs1599847663, REVEL 0.21, CADD 23.80
- L103F (p.Leu103Phe), ExAC rs775189541, TOPMed rs775189541, gnomAD rs775189541, REVEL 0.43, CADD 23.90
- S104R (p.Ser104Arg), 1000Genomes rs114540811, ExAC rs114540811, TOPMed rs114540811, gnomAD rs114540811, REVEL 0.26, CADD 18.80, Likely benign
- D105A (p.Asp105Ala), rs2513785055, ClinGen CA405410950, ClinVar RCV003040380, Likely pathogenic, not provided
- D105N (p.Asp105Asn), rs386833932, ClinGen CA250218, cosmic curated COSV62289, ClinVar RCV000049906, REVEL 0.61, CADD 25.50, Likely pathogenic, not provided; Finnish congenital nephrotic syndrome; Nephrotic syndrome
- D106E (p.Asp106Glu), ExAC rs770909581, TOPMed rs770909581, gnomAD rs770909581, REVEL 0.35, CADD 0.81, Likely benign
- D106G (p.Asp106Gly), ExAC rs776058104, gnomAD rs776058104, REVEL 0.37, CADD 25.20
- D106Y (p.Asp106Tyr), ExAC rs759088529, TOPMed rs759088529, gnomAD rs759088529, REVEL 0.46, CADD 24.70
- A107E (p.Ala107Glu), rs386833934, ClinGen CA405410912, NCI-TCGA Cosmic COSV6229, cosmic curated COSV62290, REVEL 0.46, CADD 24.50, Uncertain significance, not specified
- A107T (p.Ala107Thr), rs386833933, ClinGen CA250221, cosmic curated COSV62286, ClinVar RCV000049907, REVEL 0.40, CADD 23.00, Conflicting interpretations, not provided; Finnish congenital nephrotic syndrome; not specified
- A107V (p.Ala107Val), rs386833934, ClinGen CA250223, ClinVar RCV000049908, UniProt VAR 064196, REVEL 0.42, CADD 24.80, Uncertain significance, Finnish congenital nephrotic syndrome
- E108* (p.Glu108Ter), rs2146831931, ClinGen CA405410899, ClinVar RCV001921322, Ensembl rs2146831931, Pathogenic
- E108D (p.Glu108Asp), Ensembl rs1599847618, REVEL 0.02, CADD 12.60
- E108K (p.Glu108Lys), NCI-TCGA Cosmic COSV6229, cosmic curated COSV62290, REVEL 0.20, CADD 10.10, Variant assessed as somatic; moderate impact.
- Y109* (p.Tyr109Ter), ExAC rs779228955, TOPMed rs779228955, gnomAD rs779228955, CADD 35.00, Likely benign
- Y109C (p.Tyr109Cys), Ensembl rs993777150, REVEL 0.78, CADD 29.90, Uncertain significance, Finnish congenital nephrotic syndrome
- Y109H (p.Tyr109His), rs747849728, ClinGen CA9390847, ClinVar RCV000670152, ExAC rs747849728, REVEL 0.82, CADD 26.80, Uncertain significance, Finnish congenital nephrotic syndrome
- Y109S (p.Tyr109Ser), Ensembl rs993777150
- C111* (p.Cys111Ter), rs755089331, ClinGen CA405410805, ClinVar RCV002309441, Likely pathogenic
- Q112* (p.Gln112Ter), TOPMed rs1973251766
- Q112H (p.Gln112His), Ensembl rs1179960247
- Q112P (p.Gln112Pro), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V113I (p.Val113Ile), TOPMed rs1973251386, REVEL 0.28, CADD 23.70
- G114S (p.Gly114Ser), cosmic curated COSV62286, ExAC rs780271110, TOPMed rs780271110, gnomAD rs780271110, REVEL 0.09, CADD 5.75
- G114V (p.Gly114Val), Ensembl rs2146831868
- R115C (p.Arg115Cys), ExAC rs756755401, TOPMed rs756755401, gnomAD rs756755401, REVEL 0.27, CADD 25.80, Uncertain significance, Finnish congenital nephrotic syndrome
- R115H (p.Arg115His), ExAC rs768047120, TOPMed rs768047120, gnomAD rs768047120, REVEL 0.30, CADD 25.20, Uncertain significance
- R115L (p.Arg115Leu), rs768047120, ExAC rs768047120, TOPMed rs768047120, gnomAD rs768047120, REVEL 0.36, CADD 25.20, Uncertain significance, Finnish congenital nephrotic syndrome
Public NPHS1 analysis runs
- NPHS1 analysis run — NPHS1 (1,958 variants) — completed 2026-08-19