MMACHC (Q9Y4U1) variants and mutations
MMACHC (also known as Q9Y4U1) is a human protein-coding gene encoding a cyanocobalamin reductase / alkylcobalamin dealkylase protein. It processes intracellular cobalamin so that vitamin B12 can be converted into the active cofactors needed for methionine synthase and methylmalonyl-CoA mutase. Biallelic loss causes cblC disease, with combined methylmalonic acidemia and homocystinuria and highly variable neurologic and systemic manifestations. This analysis covers 726 MMACHC variants and mutations. Of these, 86% have computational variant effect predictions. Disease context includes Methylmalonic acidemia with homocystinuria, type cblC, methylmalonic aciduria and homocystinuria type cblC, and Methylmalonic acidemia with homocystinuria. Example MMACHC variants include M1I, M1L, and M1R.
Variant analysis overview
- Gene: MMACHC
- Protein: Q9Y4U1
- UniProt accession: Q9Y4U1
- Organism: Homo sapiens
- Variants analyzed: 726
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 457 unspecified-consequence records; 97 missense variants; 102 synonymous variants; 48 frameshift variants; 13 in-frame deletions; 4 stop-gained variants; 4 splice-region variants; 1 in-frame insertions
- Prediction scores: 624 variants have prediction scores (86% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: Methylmalonic acidemia with homocystinuria, type cblC, methylmalonic aciduria and homocystinuria type cblC, Methylmalonic acidemia with homocystinuria, hereditary disease, disorders of vitamin D metabolism, methylmalonic aciduria due to methylmalonyl-CoA mutase deficiency, Methylmalonic aciduria, Abnormality of metabolism/homeostasis, methylmalonic aciduria and homocystinuria, methylmalonic aciduria and homocystinuria type cblD, homocystinuria, atypical hemolytic-uremic syndrome.
Protein structure and variant hotspots
- Protein features: 5 binding sites; 4 post-translational modification sites.
- PTM context: 5 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable MMACHC variants
Examples include M1I, M1L, M1R, M1T, M1V, E2G, E2K, E2V. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1I (p.Met1Ile), rs779893448, ClinGen CA312724, ClinVar RCV000664762, MetaLR 0.90, MetaSVM 0.99, Pathogenic, Cobalamin C disease
- M1L (p.Met1Leu), rs758477536, ClinGen CA21825901, ClinVar RCV003497071, MetaLR 0.90, MetaSVM 0.99, Pathogenic, Cobalamin C disease
- M1R (p.Met1Arg), rs574983400, ClinGen CA340128247, ClinVar RCV000673566, MetaLR 0.92, MetaSVM 1.03, Pathogenic/Likely pathogenic, Cobalamin C disease
- M1T (p.Met1Thr), rs574983400, ClinGen CA21825904, ClinVar RCV000672157, MetaLR 0.92, MetaSVM 1.03, Uncertain significance, Cobalamin C disease
- M1V (p.Met1Val), rs758477536, ClinGen CA827593, ClinVar RCV000440436, ClinVar RCV000666093, MetaLR 0.90, MetaSVM 0.99, Pathogenic, not provided; Cobalamin C disease
- E2G (p.Glu2Gly), 1000Genomes rs543492649, ExAC rs543492649, gnomAD rs543492649
- E2K (p.Glu2Lys), TOPMed rs1454919873
- E2V (p.Glu2Val), 1000Genomes rs543492649, ExAC rs543492649, gnomAD rs543492649, REVEL 0.48, CADD 26.20
- P3R (p.Pro3Arg), rs201807738, ClinGen CA827595, ClinVar RCV002174708, ClinVar RCV002508338, REVEL 0.38, CADD 22.60, Conflicting interpretations, not provided; Cobalamin C disease
- P3A (p.Pro3Ala), gnomAD 1-45500339-C-G, REVEL 0.18, MetaLR 0.60
- P3P (p.Pro3Pro), rs199867236, gnomAD 1-45500341-G-A, CADD 8.54
- K4T (p.Lys4Thr), TOPMed rs1204198077, gnomAD rs1204198077, REVEL 0.27, CADD 2.95
- K4E (p.Lys4Glu), gnomAD 1-45500342-A-G, REVEL 0.20, MetaLR 0.65
- V5A (p.Val5Ala), ExAC rs780981680, TOPMed rs780981680, gnomAD rs780981680, Uncertain significance
- V5D (p.Val5Asp), rs780981680, ClinGen CA827596, ClinVar RCV001899154, ExAC rs780981680, REVEL 0.72, CADD 24.50, Uncertain significance, Cobalamin C disease
- A6S (p.Ala6Ser), rs747875672, NCI-TCGA Cosmic COSV6898, ExAC rs747875672, gnomAD rs747875672, REVEL 0.24, CADD 20.80, Variant assessed as somatic; moderate impact.
- A6T (p.Ala6Thr), gnomAD 1-45500348-G-A, REVEL 0.20, MetaLR 0.70
- E7K (p.Glu7Lys), rs377405910, ClinGen CA827598, ClinVar RCV001250055, ClinVar RCV006279511, REVEL 0.44, CADD 23.30, Conflicting interpretations, Cobalamin C disease; not provided
- E7S (p.Glu7Ser), rs1643516622, gnomAD 1-45500349-CA-C, CADD 22.70
- E7G (p.Glu7Gly), gnomAD 1-45500352-A-G, REVEL 0.57, MetaLR 0.77
- L8Q (p.Leu8Gln), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L8V (p.Leu8Val), gnomAD 1-45500354-C-G, REVEL 0.26, MetaLR 0.69
- Q10H (p.Gln10His), ExAC rs772838196, gnomAD rs772838196, REVEL 0.28, CADD 23.10, Uncertain significance, Cobalamin C disease
- Q10R (p.Gln10Arg), gnomAD 1-45500361-A-G, REVEL 0.20, MetaLR 0.53
- K11M (p.Lys11Met), ExAC rs748798542, gnomAD rs748798542
- K11N (p.Lys11Asn), rs770446383, ClinGen CA340128477, ClinVar RCV003277098, ExAC rs770446383, REVEL 0.26, CADD 22.70, Uncertain significance, Inborn genetic diseases
- K11del (p.Lys11del), rs2149320876, gnomAD 1-45500360-CAGA-C, CADD 22.20
- K11T (p.Lys11Thr), gnomAD 1-45500364-A-C, REVEL 0.22, MetaLR 0.65
- K11K (p.Lys11Lys), rs770446383, gnomAD 1-45500365-G-A, CADD 14.60
- I12L (p.Ile12Leu), ExAC rs773695165, gnomAD rs773695165, REVEL 0.19, CADD 19.10
- I12V (p.Ile12Val), gnomAD 1-45500366-A-G, REVEL 0.16, MetaLR 0.61
- I12I (p.Ile12Ile), gnomAD 1-45500368-C-A, CADD 14.10
- E13* (p.Glu13Ter), NCI-TCGA Cosmic COSV1012, Variant assessed as somatic; high impact.
- E13A (p.Glu13Ala), rs1010232462, ClinGen CA21825934, ClinVar RCV001863982, ClinVar RCV005601809, REVEL 0.25, CADD 23.50, Uncertain significance, not provided; Cobalamin C disease; Inborn genetic diseases
- E13K (p.Glu13Lys), ExAC rs761257132, TOPMed rs761257132, gnomAD rs761257132
- E13Q (p.Glu13Gln), ExAC rs761257132, TOPMed rs761257132, gnomAD rs761257132
- E13V (p.Glu13Val), NCI-TCGA TCGA novel, REVEL 0.35, CADD 25.30, Variant assessed as somatic; moderate impact.
- E13G (p.Glu13Gly), gnomAD 1-45500370-A-G, REVEL 0.32, MetaLR 0.74
- E13E (p.Glu13Glu), rs764626433, gnomAD 1-45500371-G-A, CADD 13.60
- D14G (p.Asp14Gly), NCI-TCGA Cosmic COSV1012, Variant assessed as somatic; moderate impact.
- D14N (p.Asp14Asn), rs563710045, ClinGen CA827605, ClinVar RCV000706168, ClinVar RCV003928175, REVEL 0.24, CADD 23.20, Conflicting interpretations, Cobalamin C disease
- D14D (p.Asp14Asp), rs141562335, gnomAD 1-45500374-C-T, CADD 14.20
- T15A (p.Thr15Ala), TOPMed rs1352943462, gnomAD rs1352943462, REVEL 0.22, CADD 17.20
- T15M (p.Thr15Met), ExAC rs765601770, gnomAD rs765601770, REVEL 0.25, CADD 21.00
- T15T (p.Thr15Thr), rs750623781, gnomAD 1-45500377-G-A, CADD 12.50
- L16P (p.Leu16Pro), TOPMed rs1299984717, gnomAD rs1299984717, REVEL 0.88, CADD 32.00, Uncertain significance, Cobalamin C disease
- L16V (p.Leu16Val), gnomAD rs1197773707, REVEL 0.73, CADD 25.50
- L16L (p.Leu16Leu), rs1366120426, gnomAD 1-45500380-A-G, CADD 14.20
- C17* (p.Cys17Ter), rs2522798223, ClinGen CA340128613, ClinVar RCV003461865, Likely pathogenic
- C17R (p.Cys17Arg), rs766500038, NCI-TCGA Cosmic COSV6898, ExAC rs766500038, gnomAD rs766500038, REVEL 0.50, CADD 23.00, Variant assessed as somatic; moderate impact.
- C17Y (p.Cys17Tyr), ExAC rs751539831, gnomAD rs751539831, REVEL 0.48, CADD 21.80
- C17S (p.Cys17Ser), rs765960386, gnomAD 1-45500378-CTA-C, CADD 29.00
- P18H (p.Pro18His), rs371004372, NCI-TCGA Cosmic COSV6898, ESP rs371004372, ExAC rs371004372, REVEL 0.55, CADD 26.60, Uncertain significance
- P18L (p.Pro18Leu), rs371004372, ClinGen CA21825952, ClinVar RCV002032102, ESP rs371004372, REVEL 0.58, CADD 27.70, Uncertain significance, Cobalamin C disease
- P18S (p.Pro18Ser), rs1323856934, ClinGen CA340128619, ClinVar RCV003486153, gnomAD rs1323856934, REVEL 0.28, CADD 22.30, Uncertain significance, Cobalamin C disease
- P18R (p.Pro18Arg), gnomAD 1-45500385-C-G, REVEL 0.62, MetaLR 0.87
- F19S (p.Phe19Ser), gnomAD rs1273105824, REVEL 0.56, CADD 26.70
- F19L (p.Phe19Leu), gnomAD 1-45500387-T-C, REVEL 0.28, MetaLR 0.57
- G20D (p.Gly20Asp), rs375909359, ClinGen CA21825955, ClinVar RCV001099136, ESP rs375909359, REVEL 0.93, CADD 29.40, Uncertain significance, Disorders of Intracellular Cobalamin Metabolism
- G20A (p.Gly20Ala), gnomAD 1-45500391-G-C, REVEL 0.93, MetaLR 0.97
- G20V (p.Gly20Val), gnomAD 1-45500391-G-T, REVEL 0.94, MetaLR 0.97
- F21L (p.Phe21Leu), gnomAD 1-45500393-T-C, REVEL 0.77, MetaLR 0.85
- E22K (p.Glu22Lys), gnomAD rs1478779847, REVEL 0.94, CADD 32.00
- E22V (p.Glu22Val), ExAC rs781106513, gnomAD rs781106513, REVEL 0.95, CADD 32.00
- E22G (p.Glu22Gly), gnomAD 1-45500397-A-G, REVEL 0.95, MetaLR 0.95
- V23F (p.Val23Phe), rs201898615, ClinGen CA827615, ClinVar RCV000308210, ClinVar RCV001700037, REVEL 0.79, CADD 23.00, Uncertain significance, not provided; Disorders of Intracellular Cobalamin Metabolism; Inborn genetic di
- V23I (p.Val23Ile), gnomAD 1-45500399-G-A, REVEL 0.29, MetaLR 0.73
- Y24* (p.Tyr24Ter), rs755881820, ClinGen CA340128765, ClinVar RCV000669100, ExAC rs755881820, Likely pathogenic
- Y24Y (p.Tyr24Tyr), rs755881820, gnomAD 1-45500404-C-T, CADD 11.60
- P25A (p.Pro25Ala), TOPMed rs1325442638, gnomAD rs1325442638, REVEL 0.70, CADD 25.40
- P25H (p.Pro25His), ExAC rs777332324, gnomAD rs777332324
- P25L (p.Pro25Leu), ExAC rs777332324, gnomAD rs777332324, REVEL 0.86, CADD 25.30
- P25T (p.Pro25Thr), TOPMed rs1325442638, gnomAD rs1325442638, REVEL 0.83, CADD 26.00
- P25P (p.Pro25Pro), rs749003802, gnomAD 1-45500407-C-A, CADD 13.30
- F26L (p.Phe26Leu), ExAC rs770431439, TOPMed rs770431439, gnomAD rs770431439, REVEL 0.80, CADD 23.90, Uncertain significance, Cobalamin C disease
- F26V (p.Phe26Val), TOPMed rs1318571220, gnomAD rs1318571220, REVEL 0.93, CADD 29.40
- F26F (p.Phe26Phe), rs770431439, gnomAD 1-45500410-C-T, CADD 16.20
- Q27R (p.Gln27Arg), rs546099787, ClinGen CA827620, ClinVar RCV000667730, UniProt VAR 024770, REVEL 0.57, CADD 25.70, Pathogenic, Cobalamin C disease
- V28A (p.Val28Ala), rs2522819806, ClinGen CA340131352, ClinVar RCV004514414, Uncertain significance, Inborn genetic diseases
- V28L (p.Val28Leu), TOPMed rs371937044, gnomAD rs371937044, REVEL 0.68, CADD 28.70
- V28M (p.Val28Met), TOPMed rs371937044, gnomAD rs371937044, REVEL 0.81, CADD 32.00
- A29S (p.Ala29Ser), TOPMed rs1643636491
- A29T (p.Ala29Thr), gnomAD 1-45507359-G-A, REVEL 0.59, CADD 24.70
- W30* (p.Trp30Ter), rs771673343, ClinGen CA827640, ClinVar RCV000671638, ExAC rs771673343, CADD 32.00, Pathogenic
- W30R (p.Trp30Arg), rs745419717, ClinGen CA827639, ClinVar RCV000685675, ExAC rs745419717, REVEL 0.94, CADD 29.60, Uncertain significance, Cobalamin C disease
- W30M (p.Trp30Met), gnomAD 1-45507359-G-GC, CADD 32.00
- W30C (p.Trp30Cys), gnomAD 1-45507364-G-C, REVEL 0.93, CADD 32.00
- Y31* (p.Tyr31Ter), rs1295015390, ClinGen CA340131374, ClinVar RCV003496556, CADD 32.00, Pathogenic
- Y31H (p.Tyr31His), gnomAD rs1400192154, REVEL 0.98, CADD 28.10
- N32N (p.Asn32Asn), gnomAD 1-45507370-T-C, CADD 10.40
- E33* (p.Glu33Ter), rs2522819881, ClinGen CA340131384, ClinVar RCV002309542, Likely pathogenic
- E33G (p.Glu33Gly), ESP rs367990231, ExAC rs367990231, TOPMed rs367990231, gnomAD rs367990231, REVEL 0.28, CADD 21.60
- E33V (p.Glu33Val), ESP rs367990231, ExAC rs367990231, TOPMed rs367990231, gnomAD rs367990231, REVEL 0.34, CADD 22.30
- E33del (p.Glu33del), gnomAD 1-45507370-TGAA-T, CADD 20.70
- L34F (p.Leu34Phe), ExAC rs758974575, gnomAD rs758974575, REVEL 0.26, CADD 19.40
- L34I (p.Leu34Ile), ExAC rs758974575, gnomAD rs758974575
- L35S (p.Leu35Ser), gnomAD 1-45507375-TCTTGC, CADD 27.60
- L35L (p.Leu35Leu), rs1415635839, gnomAD 1-45507379-G-A, CADD 9.79
- P36L (p.Pro36Leu), ExAC rs770139367, TOPMed rs770139367, gnomAD rs770139367, REVEL 0.55, CADD 23.90, Uncertain significance
- P36R (p.Pro36Arg), ExAC rs770139367, TOPMed rs770139367, gnomAD rs770139367, REVEL 0.37, CADD 21.30, Uncertain significance, Cobalamin C disease
- P36S (p.Pro36Ser), gnomAD 1-45507380-C-T, REVEL 0.26, CADD 18.70
- P37S (p.Pro37Ser), gnomAD rs1353976831, REVEL 0.36, CADD 15.00
- P37P (p.Pro37Pro), gnomAD 1-45507385-A-G, CADD 11.20
- A38T (p.Ala38Thr), gnomAD 1-45507386-G-A, REVEL 0.14, CADD 16.20
- A38A (p.Ala38Ala), rs372262322, gnomAD 1-45507388-C-T, CADD 7.16, SIFT 0.32
- F39C (p.Phe39Cys), Ensembl rs1643638931, REVEL 0.82, CADD 25.40
- F39S (p.Phe39Ser), Ensembl rs1643638931, REVEL 0.82, CADD 25.90
- F39L (p.Phe39Leu), rs1643638381, gnomAD 1-45507387-C-CA, CADD 24.40
- H40Y (p.His40Tyr), TOPMed rs933447358, REVEL 0.66, CADD 22.40
- H40L (p.His40Leu), gnomAD 1-45507393-A-T, REVEL 0.52, CADD 22.50
- H40Q (p.His40Gln), gnomAD 1-45507394-C-G, REVEL 0.23, CADD 6.38
- L41H (p.Leu41His), rs2149323197, gnomAD 1-45507395-CT-C, CADD 23.90
- P42L (p.Pro42Leu), rs763226016, ClinGen CA827645, NCI-TCGA Cosmic COSV5311, ClinVar RCV001772400, REVEL 0.31, CADD 13.30, Uncertain significance, not provided; Cobalamin C disease
- P42S (p.Pro42Ser), rs1643639134, gnomAD 1-45507396-T-TGAG, CADD 24.00
- P42A (p.Pro42Ala), gnomAD 1-45507398-C-G, REVEL 0.26, CADD 4.54
- P42P (p.Pro42Pro), rs201112314, gnomAD 1-45507400-G-A, CADD 5.08, SIFT 0.02
- L43W (p.Leu43Trp), gnomAD 1-45507392-CACCTA, CADD 25.70
- L43P (p.Leu43Pro), gnomAD 1-45507402-T-C, REVEL 0.66, CADD 24.30
- P44R (p.Pro44Arg), ExAC rs774414508, TOPMed rs774414508, gnomAD rs774414508, REVEL 0.61, CADD 23.60
- G45R (p.Gly45Arg), TOPMed rs1312343436, gnomAD rs1312343436, REVEL 0.50, CADD 23.30
- P46R (p.Pro46Arg), rs2149323209, ClinGen CA340131479, ClinVar RCV001931148, Ensembl rs2149323209, REVEL 0.41, CADD 24.10, Uncertain significance, Cobalamin C disease
- T47A (p.Thr47Ala), TOPMed rs1570829600
- T47I (p.Thr47Ile), rs200920274, ClinGen CA827649, ClinVar RCV002607810, ESP rs200920274, REVEL 0.88, CADD 24.30, Uncertain significance, Cobalamin C disease
- T47N (p.Thr47Asn), rs200920274, ClinGen CA827648, ClinVar RCV002633320, ClinVar RCV003269512, REVEL 0.83, CADD 24.00, Uncertain significance, Inborn genetic diseases; Cobalamin C disease
- T47P (p.Thr47Pro), TOPMed rs1570829600
- T47T (p.Thr47Thr), rs936938761, gnomAD 1-45507415-C-G, CADD 1.91
- L48V (p.Leu48Val), gnomAD 1-45507416-C-G, REVEL 0.81, CADD 23.20
- L48L (p.Leu48Leu), gnomAD 1-45507418-G-A, CADD 8.87
- A49P (p.Ala49Pro), rs775502093, ClinGen CA340131512, ClinVar RCV001351726, ExAC rs775502093, AlphaMissense 0.92, MetaLR 0.95, Uncertain significance, Cobalamin C disease
- A49S (p.Ala49Ser), ExAC rs775502093, TOPMed rs775502093, gnomAD rs775502093, REVEL 0.88, AlphaMissense 0.92, Uncertain significance
- A49T (p.Ala49Thr), rs775502093, ClinGen CA827650, ClinVar RCV002301124, ExAC rs775502093, REVEL 0.92, AlphaMissense 0.92, Uncertain significance, Cobalamin C disease
- A49V (p.Ala49Val), gnomAD rs1182723536, REVEL 0.87, CADD 24.50, Uncertain significance, Cobalamin C disease
- A49A (p.Ala49Ala), rs1570829648, gnomAD 1-45507421-C-T, CADD 9.47, SIFT 0.38
- F50F (p.Phe50Phe), rs760608755, gnomAD 1-45507424-C-T, CADD 7.78, SIFT 0.00
- L51M (p.Leu51Met), NCI-TCGA Cosmic COSV9942, Variant assessed as somatic; moderate impact.
- L51L (p.Leu51Leu), rs1643642147, gnomAD 1-45507427-G-C, CADD 6.10, SIFT 0.00
- V52I (p.Val52Ile), TOPMed rs1468551783, gnomAD rs1468551783, REVEL 0.52, CADD 18.30
- V52A (p.Val52Ala), gnomAD 1-45507429-T-C, REVEL 0.90, CADD 25.40
- V52V (p.Val52Val), rs763931975, gnomAD 1-45507430-A-G, CADD 8.73, SIFT 0.00
- L53F (p.Leu53Phe), rs201507059, ClinGen CA827653, ClinVar RCV003417085, 1000Genomes rs201507059, REVEL 0.76, CADD 24.30, Uncertain significance, MMACHC-related disorder
- L53P (p.Leu53Pro), rs756980496, ClinGen CA827654, ClinVar RCV000585794, ClinVar RCV003323623, REVEL 0.98, CADD 27.00, Conflicting interpretations, not specified; Cobalamin C disease
- L53V (p.Leu53Val), rs201507059, ClinGen CA21828838, ClinVar RCV003295343, 1000Genomes rs201507059, REVEL 0.55, CADD 19.50, Uncertain significance, Inborn genetic diseases
- L53L (p.Leu53Leu), rs371927733, gnomAD 1-45507433-C-T, CADD 8.71, SIFT 0.01
- S54G (p.Ser54Gly), TOPMed rs1643643021, gnomAD rs1643643021, REVEL 0.87, CADD 23.40, Uncertain significance, Cobalamin C disease
- S54N (p.Ser54Asn), gnomAD rs1173221159, REVEL 0.71, CADD 23.50
- S54R (p.Ser54Arg), rs750127773, ClinGen CA827656, ClinVar RCV001989721, ClinVar RCV004801104, REVEL 0.93, CADD 24.30, Uncertain significance, not specified; Cobalamin C disease
- S54S (p.Ser54Ser), rs750127773, gnomAD 1-45507436-C-T, CADD 10.70, SIFT 0.00
- T55M (p.Thr55Met), rs375330130, ClinGen CA827657, ClinVar RCV002681027, ClinVar RCV003481322, REVEL 0.89, CADD 24.80, Uncertain significance, Cobalamin C disease; not provided
- T55T (p.Thr55Thr), rs369883781, gnomAD 1-45507439-G-A, CADD 6.74, SIFT 0.03
- P56S (p.Pro56Ser), NCI-TCGA Cosmic COSV5311, Variant assessed as somatic; moderate impact.
- P56T (p.Pro56Thr), Ensembl rs1643643880, REVEL 0.97, CADD 24.60
- P56L (p.Pro56Leu), gnomAD 1-45507439-GC-G, CADD 26.60
- M58T (p.Met58Thr), rs756713628, ClinGen CA827660, ClinVar RCV002509971, ClinVar RCV004958562, AlphaMissense 0.66, MetaLR 0.91, Uncertain significance, Cobalamin C disease; Inborn genetic diseases; not provided
- F59L (p.Phe59Leu), ExAC rs778133848, gnomAD rs778133848, REVEL 0.98, CADD 28.10
- D60H (p.Asp60His), rs6662272, ClinGen CA292117, ClinVar RCV000126792, ClinVar RCV000224616, REVEL 0.77, CADD 26.90, Benign, Disorders of Intracellular Cobalamin Metabolism; not specified; not provided
- D60N (p.Asp60Asn), 1000Genomes rs6662272, ESP rs6662272, ExAC rs6662272, TOPMed rs6662272, REVEL 0.71, CADD 27.70, Benign
- D60D (p.Asp60Asp), rs535215325, gnomAD 1-45507454-C-T, CADD 8.90
- R61P (p.Arg61Pro), rs201777449, ClinGen CA340131703, ClinVar RCV001059924, ClinVar RCV002254949, REVEL 0.45, CADD 6.57, Pathogenic/Likely pathogenic, Cobalamin C disease; not provided
- R61Q (p.Arg61Gln), rs201777449, ClinGen CA827662, ClinVar RCV000641153, ClinVar RCV002252187, REVEL 0.23, CADD 0.28, Uncertain significance, Cobalamin C disease; See cases
- R61W (p.Arg61Trp), rs200483477, ClinGen CA312726, cosmic curated COSV53114, ClinVar RCV000186023, REVEL 0.33, CADD 24.20, Conflicting interpretations, Methylmalonic aciduria, type cblc; Inborn genetic diseases; Disorders of Intrace
- R61G (p.Arg61Gly), gnomAD 1-45507455-C-G, REVEL 0.25, CADD 22.00
- A62T (p.Ala62Thr), Ensembl rs1570829811, REVEL 0.74, CADD 22.80
- A62D (p.Ala62Asp), gnomAD 1-45507459-C-A, REVEL 0.94, CADD 25.50
- A62V (p.Ala62Val), gnomAD 1-45507459-C-T, REVEL 0.85, CADD 25.10
- L63S (p.Leu63Ser), rs1343936481, gnomAD 1-45507458-GC-G, CADD 26.90
- L63L (p.Leu63Leu), rs1643644883, gnomAD 1-45507463-C-G, CADD 8.30
- K64N (p.Lys64Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- K64S (p.Lys64Ser), rs1205537581, gnomAD 1-45507463-CA-C, CADD 28.30
- P65P (p.Pro65Pro), gnomAD 1-45507469-C-T, CADD 8.58
- F66L (p.Phe66Leu), gnomAD 1-45507472-C-G, REVEL 0.78, CADD 24.20
- L67L (p.Leu67Leu), rs1272042617, gnomAD 1-45507473-T-C, CADD 10.70
- Q68* (p.Gln68Ter), rs1570829862, ClinGen CA340131805, ClinVar RCV001004151, Ensembl rs1570829862, Likely pathogenic
- Q68H (p.Gln68His), gnomAD 1-45507478-G-C, REVEL 0.26, CADD 20.60
- S69N (p.Ser69Asn), 1000Genomes rs568459545, TOPMed rs568459545, REVEL 0.24, CADD 18.40
- S69R (p.Ser69Arg), gnomAD rs1643645633
- C70Y (p.Cys70Tyr), gnomAD 1-45507483-G-A, REVEL 0.30, CADD 7.02
- H71H (p.His71His), rs746112343, gnomAD 1-45507487-C-T, CADD 2.77
- R73* (p.Arg73Ter), rs796051995, ClinGen CA312728, ClinVar RCV000186024, ClinVar RCV000671572, CADD 32.00, Pathogenic
- R73Q (p.Arg73Gln), Ensembl rs1553162783, REVEL 0.32, CADD 0.13
- M74I (p.Met74Ile), rs772225967, ClinGen CA827667, ClinVar RCV001973606, ExAC rs772225967, REVEL 0.24, CADD 1.54, Uncertain significance, not provided; Inborn genetic diseases; Cobalamin C disease
Public MMACHC analysis runs
- MMACHC analysis run — MMACHC (726 variants) — completed 2026-08-19