KCNJ11 (Q14654) variants and mutations
KCNJ11 (also known as Q14654) is a human protein-coding gene encoding an ATP-sensitive inward rectifier potassium channel 11 protein. Together with SUR1, its ATP-sensitive potassium conductance couples pancreatic beta-cell metabolism to membrane depolarization and insulin secretion. Activating variants cause neonatal diabetes, whereas loss-of-function variants can cause congenital hyperinsulinism. This analysis covers 897 KCNJ11 variants and mutations. Of these, 86% have computational variant effect predictions. Disease context includes type 2 diabetes mellitus, hyperinsulinemic hypoglycemia, familial, 2, and diabetes mellitus, permanent neonatal 2. Example KCNJ11 variants include M1?, L2P, and L2L.
Variant analysis overview
- Gene: KCNJ11
- Protein: Q14654
- UniProt accession: Q14654
- Organism: Homo sapiens
- Variants analyzed: 897
- Variant scope: all variants
- Completed: 2026-08-18
Variant and mutation evidence
- Variant composition: 496 unspecified-consequence records; 1 stop retained variant; 2 stop lost; 194 synonymous variants; 165 missense variants; 4 in-frame deletions; 22 frameshift variants; 1 in-frame insertions; 4 stop-gained variants; 8 substitution
- Prediction scores: 771 variants have prediction scores (86% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: type 2 diabetes mellitus, hyperinsulinemic hypoglycemia, familial, 2, diabetes mellitus, permanent neonatal 2, diabetes mellitus, transient neonatal, 3, diabetes mellitus, permanent neonatal diabetes mellitus, transient neonatal diabetes mellitus, MODY, autosomal dominant hyperinsulinism due to Kir6.2 deficiency, diazoxide-resistant focal hyperinsulinism due to Kir6.2 deficiency, permanent neonatal diabetes mellitus 1, familial hyperinsulinism.
Protein structure and variant hotspots
- Protein features: 2 transmembrane segments; 6 binding sites; 2 post-translational modification sites.
- Structural context: 101 variants have structural context.
- PTM context: 4 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable KCNJ11 variants
Examples include M1?, L2P, L2L, L2M, S3C, S3F, S3Y, R4C. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1?, NCI-TCGA Cosmic COSV5685, Variant assessed as somatic; high impact.
- L2P (p.Leu2Pro), rs193922565, ClinGen CA214112, ClinVar RCV000030105, ClinVar RCV002226660, AlphaMissense 0.33, MetaLR 0.81, Conflicting interpretations, Maturity-onset diabetes of the young; Neonatal diabetes mellitus
- L2L (p.Leu2Leu), gnomAD 11-17388088-G-A, CADD 11.90
- L2M (p.Leu2Met), gnomAD 11-17388088-G-T, REVEL 0.41, CADD 25.00
- S3C (p.Ser3Cys), rs587783674, ClinGen CA172350, ClinVar RCV000146121, Ensembl rs587783674, AlphaMissense 0.49, MetaLR 0.60, Pathogenic, Neonatal insulin-dependent diabetes mellitus
- S3F (p.Ser3Phe), rs587783674, ClinGen CA379777902, ClinVar RCV002226805, Ensembl rs587783674, AlphaMissense 0.49, MetaLR 0.60, Uncertain significance, Type 2 diabetes mellitus
- S3Y (p.Ser3Tyr), gnomAD 11-17388084-G-T, REVEL 0.46, CADD 28.20
- R4C (p.Arg4Cys), rs543286136, ClinGen CA5902349, NCI-TCGA Cosmic COSV1002, ClinVar RCV001277856, REVEL 0.78, CADD 32.00, Uncertain significance, Type 2 diabetes mellitus; Diabetes mellitus, transient neonatal, 3; Hyperinsulin
- R4H (p.Arg4His), rs769283457, ClinGen CA5902348, NCI-TCGA Cosmic COSV5684, ClinVar RCV003236448, REVEL 0.76, CADD 28.70, Uncertain significance, not specified
- R4L (p.Arg4Leu), NCI-TCGA Cosmic COSV5684, Variant assessed as somatic; moderate impact.
- R4S (p.Arg4Ser), rs543286136, ClinGen CA238613, ClinVar RCV000173148, 1000Genomes rs543286136, REVEL 0.74, CADD 32.00, Uncertain significance, not provided
- K5N (p.Lys5Asn), TOPMed rs1953594307
- G6D (p.Gly6Asp), TOPMed rs1388209372, gnomAD rs1388209372, REVEL 0.59, CADD 26.00, Uncertain significance, not provided
- G6S (p.Gly6Ser), gnomAD rs1325935600, REVEL 0.33, CADD 21.80
- G6V (p.Gly6Val), gnomAD 11-17388075-C-A, REVEL 0.62, CADD 26.50
- G6C (p.Gly6Cys), gnomAD 11-17388076-C-A, REVEL 0.65, CADD 27.20
- I7S (p.Ile7Ser), gnomAD rs1390974211, REVEL 0.59, CADD 28.70
- I7V (p.Ile7Val), gnomAD 11-17388073-T-C, REVEL 0.30, CADD 23.10
- I8I (p.Ile8Ile), rs1228103724, gnomAD 11-17388068-G-A, CADD 11.00
- I8V (p.Ile8Val), gnomAD 11-17388070-T-C, REVEL 0.37, CADD 21.40
- I8F (p.Ile8Phe), gnomAD 11-17388070-T-A, REVEL 0.59, CADD 25.70
- P9H (p.Pro9His), Ensembl rs1953594033, Uncertain significance, Permanent neonatal diabetes mellitus
- P9L (p.Pro9Leu), rs1953594033, ClinGen CA379777721, NCI-TCGA Cosmic COSV1002, ClinVar RCV002821529, AlphaMissense 0.41, MetaLR 0.75, Uncertain significance, Inborn genetic diseases
- P9P (p.Pro9Pro), gnomAD 11-17388065-G-T, CADD 1.42
- E10K (p.Glu10Lys), rs587783667, ClinGen CA172324, ClinVar RCV000146105, ClinVar RCV002227073, REVEL 0.62, AlphaMissense 0.24, Conflicting interpretations, not specified; Maturity-onset diabetes of the young
- E10Q (p.Glu10Gln), rs587783667, ClinGen CA379777702, ClinVar RCV000986133, gnomAD rs587783667, AlphaMissense 0.24, MetaLR 0.71, Likely benign, not provided
- E10E (p.Glu10Glu), rs2133381087, gnomAD 11-17388062-C-T, CADD 10.90
- E10D (p.Glu10Asp), gnomAD 11-17388062-C-G, REVEL 0.27, CADD 16.60
- E11* (p.Glu11Ter), rs542961309, ClinGen CA379777663, ClinVar RCV003573151, AlphaMissense 0.29, MetaLR 0.59, Pathogenic
- E11K (p.Glu11Lys), TOPMed rs542961309, gnomAD rs542961309, REVEL 0.52, AlphaMissense 0.29
- E11E (p.Glu11Glu), rs2133381079, gnomAD 11-17388059-T-C, CADD 12.30
- Y12* (p.Tyr12Ter), rs104894236, ClinGen CA254517, ClinVar RCV000009208, ClinVar RCV001851756, CADD 27.60, Pathogenic
- Y12Y (p.Tyr12Tyr), rs104894236, gnomAD 11-17388056-G-A, CADD 1.81
- V13M (p.Val13Met), rs139079635, ClinGen CA5902345, ClinVar RCV002072596, ClinVar RCV002552365, REVEL 0.32, CADD 19.80, Conflicting interpretations, not specified; Inborn genetic diseases; not provided
- V13V (p.Val13Val), rs1231032422, gnomAD 11-17388053-C-T, CADD 12.60
- L14R (p.Leu14Arg), NCI-TCGA Cosmic COSV1002, Variant assessed as somatic; moderate impact.
- T15I (p.Thr15Ile), rs1200722713, gnomAD rs1200722713, REVEL 0.44, CADD 25.60, Variant assessed as somatic; moderate impact.
- T15T (p.Thr15Thr), rs746264957, gnomAD 11-17388047-T-A, CADD 2.06
- R16C (p.Arg16Cys), ExAC rs778405781, TOPMed rs778405781, gnomAD rs778405781, REVEL 0.63, CADD 28.40, Uncertain significance, Diabetes mellitus, transient neonatal, 3; Hyperinsulinemic hypoglycemia, familia
- R16H (p.Arg16His), rs770609243, ClinGen CA5902342, ClinVar RCV000509563, ClinVar RCV002226712, REVEL 0.52, CADD 24.50, Uncertain significance, Type 2 diabetes mellitus; Diabetes mellitus, transient neonatal, 3; Hyperinsulin
- R16S (p.Arg16Ser), gnomAD 11-17388046-G-T, REVEL 0.40, CADD 23.70
- L17L (p.Leu17Leu), gnomAD 11-17388041-C-T, CADD 3.88
- L17M (p.Leu17Met), gnomAD 11-17388043-G-T, REVEL 0.41, CADD 23.90
- A18E (p.Ala18Glu), rs41309072, ClinGen CA379777497, ClinVar RCV002295865, AlphaMissense 0.16, MetaLR 0.21, Uncertain significance, not provided
- A18G (p.Ala18Gly), rs41309072, UniProt VAR 055978, Ensembl rs41309072, AlphaMissense 0.16, MetaLR 0.21
- A18T (p.Ala18Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A18A (p.Ala18Ala), rs193922564, gnomAD 11-17388038-T-C, CADD 3.37
- E19G (p.Glu19Gly), Ensembl rs2133381035
- E19Q (p.Glu19Gln), NCI-TCGA Cosmic COSV5684, Variant assessed as somatic; moderate impact.
- E19E (p.Glu19Glu), rs748791717, gnomAD 11-17388035-C-T, CADD 8.82
- D20A (p.Asp20Ala), Ensembl rs1591696371
- D20E (p.Asp20Glu), TOPMed rs1953593177, Uncertain significance, not specified
- D20D (p.Asp20Asp), gnomAD 11-17388032-G-A, CADD 9.34
- D20N (p.Asp20Asn), gnomAD 11-17388034-C-T, REVEL 0.26, CADD 22.90
- P21L (p.Pro21Leu), Ensembl rs1953593069, REVEL 0.42, CADD 21.40, Conflicting interpretations, Diabetes mellitus, transient neonatal, 3; Hyperinsulinemic hypoglycemia, familia
- P21S (p.Pro21Ser), NCI-TCGA TCGA novel, REVEL 0.44, CADD 18.90, Variant assessed as somatic; moderate impact.
- P21T (p.Pro21Thr), rs1393796559, ClinGen CA379777433, ClinVar RCV003336590, ClinVar RCV005047539, REVEL 0.44, CADD 19.10, Uncertain significance, Type 1 diabetes mellitus 20; Type 2 diabetes mellitus; Diabetes mellitus type 1
- A22T (p.Ala22Thr), TOPMed rs1953593027, Uncertain significance, Inborn genetic diseases
- A22A (p.Ala22Ala), gnomAD 11-17388026-G-T, CADD 0.65
- A22V (p.Ala22Val), gnomAD 11-17388027-G-A, REVEL 0.16, CADD 16.90
- A22P (p.Ala22Pro), gnomAD 11-17388028-C-CAG, CADD 18.30
- K23* (p.Lys23Ter), 1000Genomes rs5219, ESP rs5219, ExAC rs5219, TOPMed rs5219, Benign
- K23E (p.Lys23Glu), rs5219, ClinGen CA119831, ClinVar RCV000009214, ClinVar RCV000020356, REVEL 0.17, CADD 20.30, Likely benign, Diabetes mellitus, transient neonatal, 3; Type 2 diabetes mellitus; Maturity-ons
- K23Q (p.Lys23Gln), 1000Genomes rs5219, ESP rs5219, ExAC rs5219, TOPMed rs5219, Benign
- K23N (p.Lys23Asn), gnomAD 11-17388023-C-A, REVEL 0.21, CADD 19.00
- K23R (p.Lys23Arg), gnomAD 11-17388024-T-C, REVEL 0.24, CADD 21.80
- P24S (p.Pro24Ser), gnomAD rs1331359127, REVEL 0.33, CADD 21.20
- P24R (p.Pro24Arg), gnomAD 11-17388021-G-C, REVEL 0.49, CADD 25.70
- R27C (p.Arg27Cys), rs752507753, ClinGen CA277131, ClinVar RCV000193401, ClinVar RCV001277854, REVEL 0.49, CADD 27.30, Uncertain significance, Maturity-onset diabetes of the young; not provided
- R27H (p.Arg27His), rs774714794, ClinGen CA5902339, ClinVar RCV000389894, ClinVar RCV001833339, REVEL 0.15, CADD 13.20, Conflicting interpretations, not specified; Maturity-onset diabetes of the young; Maturity-onset diabetes of
- R27P (p.Arg27Pro), ExAC rs774714794, TOPMed rs774714794, gnomAD rs774714794, Benign
- A28G (p.Ala28Gly), ExAC rs754683593, TOPMed rs754683593, gnomAD rs754683593, REVEL 0.26, CADD 18.80, Uncertain significance
- A28V (p.Ala28Val), rs754683593, ClinGen CA5902338, ClinVar RCV001375994, ClinVar RCV005050360, REVEL 0.24, CADD 19.80, Uncertain significance, Diabetes mellitus, transient neonatal, 3; Type 2 diabetes mellitus; Maturity-ons
- R29C (p.Arg29Cys), rs751424820, NCI-TCGA Cosmic COSV5685, ExAC rs751424820, TOPMed rs751424820, REVEL 0.45, CADD 25.30, Variant assessed as somatic; moderate impact.
- R29H (p.Arg29His), rs988002138, ClinGen CA218400191, ClinVar RCV001757910, ClinVar RCV005040346, REVEL 0.34, CADD 22.80, Uncertain significance, not provided; Diabetes mellitus, transient neonatal, 3; Type 2 diabetes mellitus
- R29R (p.Arg29Arg), rs539327013, gnomAD 11-17388005-G-C, CADD 0.15
- R31L (p.Arg31Leu), 1000Genomes rs571564577, ExAC rs571564577, TOPMed rs571564577, gnomAD rs571564577, REVEL 0.42, CADD 19.60
- R31Q (p.Arg31Gln), 1000Genomes rs571564577, ExAC rs571564577, TOPMed rs571564577, gnomAD rs571564577, REVEL 0.33, CADD 18.90, Uncertain significance, not provided
- R31W (p.Arg31Trp), rs757621300, ClinGen CA5902335, ClinVar RCV001105581, ClinVar RCV001105582, REVEL 0.51, CADD 23.00, Uncertain significance, Maturity-onset diabetes of the young type 13; Diabetes mellitus, transient neona
- R31R (p.Arg31Arg), rs1377294667, gnomAD 11-17387999-C-T, CADD 7.95
- R32R (p.Arg32Arg), gnomAD 11-17387996-C-T, CADD 10.60
- R32K (p.Arg32Lys), gnomAD 11-17387997-C-T, REVEL 0.29, CADD 14.10
- A33D (p.Ala33Asp), Ensembl rs1591696296
- A33A (p.Ala33Ala), rs1489389760, gnomAD 11-17387993-G-A, CADD 10.10
- A33P (p.Ala33Pro), rs1197452068, gnomAD 11-17387994-GC-G, CADD 27.30
- A33V (p.Ala33Val), gnomAD 11-17387994-G-A, REVEL 0.55, CADD 24.50
- A33S (p.Ala33Ser), gnomAD 11-17387995-C-A, REVEL 0.52, CADD 22.80
- R34C (p.Arg34Cys), rs954727530, ClinGen CA218400169, ClinVar RCV001855597, ClinVar RCV002225111, REVEL 0.94, CADD 31.00, Pathogenic/Likely pathogenic, Familial hyperinsulinism; Monogenic diabetes; Permanent neonatal diabetes mellit
- R34G (p.Arg34Gly), TOPMed rs954727530, gnomAD rs954727530, REVEL 0.93, CADD 28.20, Likely pathogenic, Hyperinsulinemic hypoglycemia, familial, 2
- R34H (p.Arg34His), rs141145502, ClinGen CA218400168, ClinVar RCV001588331, ClinVar RCV001832822, REVEL 0.96, CADD 27.70, Pathogenic/Likely pathogenic, Hyperinsulinemic hypoglycemia, familial, 2; Permanent neonatal diabetes mellitus
- R34L (p.Arg34Leu), ESP rs141145502, ExAC rs141145502, TOPMed rs141145502, gnomAD rs141145502, REVEL 0.96, CADD 27.30, Pathogenic, in HHF2
- F35L (p.Phe35Leu), rs193929333, ClinGen CA341714, ClinVar RCV000020345, ClinVar RCV002226651, AlphaMissense 0.93, MetaLR 0.73, Benign, Neonatal hypoglycemia
- F35S (p.Phe35Ser), Ensembl rs41314517
- F35V (p.Phe35Val), rs193929333, ClinGen CA341716, ClinVar RCV000020346, UniProt VAR 026499, AlphaMissense 0.93, MetaLR 0.73, not provided, Permanent neonatal diabetes mellitus
- V36V (p.Val36Val), rs112070496, gnomAD 11-17387984-C-T, CADD 11.30
- V36A (p.Val36Ala), gnomAD 11-17387985-A-G, REVEL 0.94, CADD 26.20
- V36E (p.Val36Glu), gnomAD 11-17387985-A-T, REVEL 0.97, CADD 27.50
- S37C (p.Ser37Cys), gnomAD rs1375461209, REVEL 0.60, CADD 25.90, Uncertain significance, Diabetes mellitus, transient neonatal, 3; Hyperinsulinemic hypoglycemia, familia
- S37Y (p.Ser37Tyr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S37S (p.Ser37Ser), gnomAD 11-17387981-G-A, CADD 13.00
- S37F (p.Ser37Phe), gnomAD 11-17387982-G-A, REVEL 0.46, CADD 24.30
- K38E (p.Lys38Glu), rs2496412209, ClinGen CA379776881, ClinVar RCV003228205, ClinVar RCV005414682, Conflicting interpretations, not provided; Hyperinsulinemic hypoglycemia, familial, 2
- K38R (p.Lys38Arg), gnomAD 11-17387979-T-C, REVEL 0.90, CADD 26.90
- K38Q (p.Lys38Gln), gnomAD 11-17387980-T-G, REVEL 0.91, CADD 26.60
- G40D (p.Gly40Asp), rs1001873841, ClinGen CA218400149, ClinVar RCV002227198, ClinVar RCV003558487, REVEL 0.99, CADD 26.80, Conflicting interpretations, Familial hyperinsulinism; Diabetes mellitus, transient neonatal, 3; Type 2 diabe
- G40S (p.Gly40Ser), Ensembl rs1564865782
- N41H (p.Asn41His), gnomAD rs1311750275, REVEL 0.33, CADD 22.80
- N41N (p.Asn41Asn), gnomAD 11-17387969-G-A, CADD 9.98
- N41T (p.Asn41Thr), gnomAD 11-17387970-T-G, REVEL 0.27, CADD 22.60
- C42F (p.Cys42Phe), 1000Genomes rs534808921, ExAC rs534808921, gnomAD rs534808921, REVEL 0.96, CADD 26.80
- C42R (p.Cys42Arg), rs80356610, ClinGen CA119829, ClinVar RCV000009211, ClinVar RCV000020347, AlphaMissense 0.97, MetaLR 0.85, Conflicting interpretations, Maturity-onset diabetes of the young; not provided
- C42Y (p.Cys42Tyr), 1000Genomes rs534808921, ExAC rs534808921, gnomAD rs534808921
- N43K (p.Asn43Lys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- N43N (p.Asn43Asn), rs1344671029, gnomAD 11-17387963-G-A, CADD 8.67
- N43S (p.Asn43Ser), gnomAD 11-17387964-T-C, REVEL 0.84, CADD 24.00
- V44A (p.Val44Ala), rs2496412079, ClinGen CA379776612, ClinVar RCV003574145, Likely pathogenic, not provided
- V44M (p.Val44Met), rs1282255458, ClinGen CA379776641, ClinVar RCV001817931, ClinVar RCV003772341, REVEL 0.87, CADD 25.50, Conflicting interpretations, not provided; Hyperinsulinemic hypoglycemia, familial, 2; not specified
- V44V (p.Val44Val), gnomAD 11-17387960-C-T, CADD 8.57
- A45S (p.Ala45Ser), gnomAD 11-17387959-C-A, REVEL 0.60, CADD 23.50
- H46Y (p.His46Tyr), UniProt VAR 031332, Pathogenic, not provided
- H46H (p.His46His), gnomAD 11-17387954-G-A, CADD 11.10
- K47E (p.Lys47Glu), gnomAD 11-17387953-T-C, REVEL 0.71, CADD 25.30
- I49M (p.Ile49Met), ExAC rs768117265, TOPMed rs768117265, Uncertain significance, not provided; Inborn genetic diseases
- I49V (p.Ile49Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R50G (p.Arg50Gly), rs1221366142, ClinGen CA379776373, ClinVar RCV003062336, AlphaMissense 0.44, MetaLR 0.94, Pathogenic, not provided
- R50L (p.Arg50Leu), rs80356611, ClinGen CA379776349, ClinVar RCV002227391, Ensembl rs80356611, REVEL 0.84, AlphaMissense 0.56, Likely risk allele, Transitory neonatal diabetes mellitus
- R50P (p.Arg50Pro), rs80356611, ClinGen CA340803, ClinVar RCV000009205, ClinVar RCV001089464, AlphaMissense 0.56, MetaLR 0.83, Pathogenic, KCNJ11-related disorder
- R50Q (p.Arg50Gln), rs80356611, ClinGen CA214108, ClinVar RCV000030103, ClinVar RCV000518206, AlphaMissense 0.56, MetaLR 0.83, Pathogenic/Likely pathogenic, Diabetes; not provided; Neonatal diabetes mellitus
- R50W (p.Arg50Trp), rs1221366142, ClinGen CA379776370, ClinVar RCV003740019, TOPMed rs1221366142, REVEL 0.91, AlphaMissense 0.44, Conflicting interpretations, not provided
- R50R (p.Arg50Arg), rs1221397837, gnomAD 11-17387942-C-T, CADD 5.71
- E51* (p.Glu51Ter), rs2496412015, ClinGen CA379776316, ClinVar RCV003557566, CADD 37.00, Pathogenic
- E51A (p.Glu51Ala), rs1953591118, gnomAD 11-17387933-GCCCT, CADD 32.00
- E51E (p.Glu51Glu), gnomAD 11-17387939-C-T, CADD 11.80
- E51S (p.Glu51Ser), rs1313986273, gnomAD 11-17387940-TC-T, CADD 29.90
- E51K (p.Glu51Lys), gnomAD 11-17387941-C-T, REVEL 0.79, CADD 25.20
- Q52* (p.Gln52Ter), rs879253757, ClinGen CA10584023, ClinVar RCV000234886, ClinVar RCV002226700, CADD 38.00, Pathogenic, in PNDM2
- Q52R (p.Gln52Arg), rs193929337, ClinGen CA341718, ClinVar RCV000020348, ClinVar RCV002227044, AlphaMissense 0.30, MetaLR 0.19, Benign, Transitory neonatal diabetes mellitus
- G53D (p.Gly53Asp), rs80356615, ClinGen CA119837, ClinVar RCV000009222, ClinVar RCV000020349, AlphaMissense 0.86, MetaLR 0.90, Benign, Neonatal hypoglycemia
- G53R (p.Gly53Arg), rs80356613, ClinGen CA340811, ClinVar RCV000009219, UniProt VAR 026502, AlphaMissense 0.47, MetaLR 0.83, Pathogenic, Diabetes mellitus, transient neonatal, 3
- G53S (p.Gly53Ser), rs80356613, ClinGen CA340809, ClinVar RCV000009218, ClinVar RCV002226644, REVEL 0.79, AlphaMissense 0.47, Conflicting interpretations, Transitory neonatal diabetes mellitus; Maturity-onset diabetes of the young; Typ
- G53G (p.Gly53Gly), gnomAD 11-17387933-G-A, CADD 12.50
- R54C (p.Arg54Cys), rs375848765, ClinGen CA5902330, ClinVar RCV000516616, ClinVar RCV002227174, REVEL 0.93, CADD 32.00, Conflicting interpretations, not specified; not provided; Maturity-onset diabetes of the young
- R54H (p.Arg54His), rs587783666, ClinGen CA271562, ClinVar RCV000146103, ClinVar RCV002227072, REVEL 0.96, CADD 28.70, Conflicting interpretations, Hyperinsulinemic hypoglycemia; Hyperinsulinemic hypoglycemia, familial, 2; not p
- R54P (p.Arg54Pro), gnomAD 11-17387931-C-CG, CADD 32.00
- R54G (p.Arg54Gly), gnomAD 11-17387932-G-C, REVEL 0.96, CADD 29.40
- F55L (p.Phe55Leu), rs1343400778, ClinGen CA379776138, ClinVar RCV003062335, ClinVar RCV003459722, REVEL 0.92, CADD 25.10, Conflicting interpretations, not provided; Type 2 diabetes mellitus
- L56L (p.Leu56Leu), rs1336022547, gnomAD 11-17387924-C-A, CADD 8.05
- L56V (p.Leu56Val), gnomAD 11-17387926-G-C, REVEL 0.83, CADD 25.60
- Q57K (p.Gln57Lys), gnomAD rs1953590851, REVEL 0.71, CADD 24.70
- Q57H (p.Gln57His), gnomAD 11-17387921-C-A, REVEL 0.74, CADD 24.60
- Q57L (p.Gln57Leu), gnomAD 11-17387922-T-A, REVEL 0.61, CADD 23.20
- Q57E (p.Gln57Glu), gnomAD 11-17387923-G-C, REVEL 0.71, CADD 24.30
- D58E (p.Asp58Glu), rs1237212288, ClinGen CA379776022, ClinVar RCV000517720, TOPMed rs1237212288, AlphaMissense 1.00, MetaLR 0.51, Uncertain significance, not provided
- D58H (p.Asp58His), NCI-TCGA Cosmic COSV5684, Variant assessed as somatic; moderate impact.
- D58D (p.Asp58Asp), rs1237212288, gnomAD 11-17387918-G-A, AlphaMissense 1.00, MetaLR 0.51
- D58A (p.Asp58Ala), gnomAD 11-17387919-T-G, REVEL 0.99, CADD 30.00
- V59G (p.Val59Gly), rs80356617, ClinGen CA119827, ClinVar RCV000009204, ClinVar RCV000020350, AlphaMissense 0.76, MetaLR 0.86, Likely benign, Transitory neonatal diabetes mellitus
- V59M (p.Val59Met), rs80356616, ClinGen CA119823, ClinVar RCV000009201, ClinVar RCV000030665, REVEL 0.77, CADD 24.10, Pathogenic, Diabetes mellitus, permanent neonatal 2; not provided; Neonatal diabetes mellitu
- F60L (p.Phe60Leu), ExAC rs770553801, gnomAD rs770553801, REVEL 0.97, CADD 29.50
- F60S (p.Phe60Ser), rs387906783, ClinGen CA379775970, ClinVar RCV000500789, Ensembl rs387906783, AlphaMissense 0.98, MetaLR 0.46, Uncertain significance, not specified
- F60Y (p.Phe60Tyr), rs387906783, ClinGen CA128966, ClinVar RCV000023046, ClinVar RCV002226654, AlphaMissense 0.98, MetaLR 0.46, Uncertain significance, Hyperinsulinemia
- F60F (p.Phe60Phe), gnomAD 11-17387912-G-A, CADD 12.10
- T62M (p.Thr62Met), rs1057518775, ClinGen CA379775836, ClinVar RCV000500297, ClinVar RCV002227172, REVEL 0.95, AlphaMissense 0.89, Conflicting interpretations, Maturity-onset diabetes of the young; not specified; not provided
- T62R (p.Thr62Arg), rs1057518775, ClinGen CA16043457, ClinVar RCV000415398, gnomAD rs1057518775, AlphaMissense 0.89, MetaLR 0.95, Likely pathogenic, Hyperinsulinemia; Atopic eczema; Hypoglycemia
- T62T (p.Thr62Thr), rs748877741, gnomAD 11-17387906-C-T, CADD 4.21
- L63M (p.Leu63Met), gnomAD rs1953590561, REVEL 0.68, CADD 23.80
- L63V (p.Leu63Val), gnomAD rs1953590561
- L63L (p.Leu63Leu), rs1173987170, gnomAD 11-17387903-C-A, CADD 9.19
- V64L (p.Val64Leu), rs115716690, UniProt VAR 073682, 1000Genomes rs115716690, ESP rs115716690, REVEL 0.92, AlphaMissense 0.93, Uncertain significance, Diabetes mellitus, transient neonatal, 3; Hyperinsulinemic hypoglycemia, familia
- V64M (p.Val64Met), rs115716690, ClinGen CA379775801, ClinVar RCV002052018, 1000Genomes rs115716690, AlphaMissense 0.93, MetaLR 0.41, Likely pathogenic, Neonatal diabetes mellitus; DEND syndrome
- V64V (p.Val64Val), rs769251241, gnomAD 11-17387900-C-T, CADD 11.20
- D65D (p.Asp65Asp), rs1488482081, gnomAD 11-17387897-G-A, CADD 11.30
- L66F (p.Leu66Phe), Ensembl rs771238609
- K67N (p.Lys67Asn), rs747719667, UniProt VAR 026506, ExAC rs747719667, gnomAD rs747719667, REVEL 0.81, CADD 23.80, Pathogenic, in HHF2
- W68G (p.Trp68Gly), gnomAD rs1474444717, REVEL 0.99, CADD 32.00
- W68* (p.Trp68Ter), gnomAD 11-17387889-C-T, CADD 37.00
- P69S (p.Pro69Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P69T (p.Pro69Thr), ESP rs372565142, ExAC rs372565142, TOPMed rs372565142, gnomAD rs372565142, REVEL 0.52, CADD 23.60
- H70Q (p.His70Gln), Ensembl rs749829780, REVEL 0.77, CADD 25.20
- H70H (p.His70His), gnomAD 11-17387882-G-A, CADD 10.40
Public KCNJ11 analysis runs
- KCNJ11 analysis run — KCNJ11 (897 variants) — completed 2026-08-18