ERCC2 (P18074) variants and mutations
ERCC2 (also known as P18074) is a human protein-coding gene encoding a general transcription and DNA repair factor IIH helicase subunit XPD protein. Its XPD helicase activity unwinds damaged DNA during nucleotide-excision repair and also supports transcription initiation within TFIIH. Biallelic pathogenic variants cause xeroderma pigmentosum, trichothiodystrophy, or combined DNA-repair syndromes depending on the functional defect. This analysis covers 1,693 ERCC2 variants and mutations. Of these, 72% have computational variant effect predictions. Disease context includes trichothiodystrophy 1, photosensitive, cerebrooculofacioskeletal syndrome 2, and Xeroderma pigmentosum complementation group D. Example ERCC2 variants include M1T, M1V, and K2N.
Variant analysis overview
- Gene: ERCC2
- Protein: P18074
- UniProt accession: P18074
- Organism: Homo sapiens
- Variants analyzed: 1693
- Variant scope: all variants
- Completed: 2026-08-18
Variant and mutation evidence
- Variant composition: 1,481 unspecified-consequence records; 2 stop lost; 57 synonymous variants; 19 frameshift variants; 102 missense variants; 16 in-frame deletions; 1 protein altering variant; 6 in-frame insertions; 2 splice-region variants; 2 stop-gained variants; 4 substitution
- Prediction scores: 1,222 variants have prediction scores (72% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: trichothiodystrophy 1, photosensitive, cerebrooculofacioskeletal syndrome 2, Xeroderma pigmentosum complementation group D, xeroderma pigmentosum group D, trichothiodystrophy, xeroderma pigmentosum, xeroderma pigmentosum-Cockayne syndrome complex, urinary bladder cancer, COFS syndrome, photosensitive trichothiodystrophy, HIV infectious disease, urinary bladder carcinoma.
Protein structure and variant hotspots
- Protein features: 1 domains; 5 binding sites.
- Structural context: 541 variants have structural context.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable ERCC2 variants
Examples include M1T, M1V, K2N, N4K, V5L, D6G, D6N, G7W. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1T (p.Met1Thr), rs764073718, ClinGen CA9513993, ClinVar RCV002042671, MetaLR 0.52, MetaSVM -0.03, Uncertain significance, not provided
- M1V (p.Met1Val), rs757252017, ClinGen CA9513995, ClinVar RCV002240084, ClinVar RCV003093916, MetaLR 0.45, MetaSVM -0.32, Uncertain significance, not specified; not provided
- K2N (p.Lys2Asn), rs200443634, ClinGen CA9513959, ClinVar RCV003053010, ClinVar RCV003170998, REVEL 0.42, CADD 26.50, Uncertain significance, not provided; Inborn genetic diseases
- N4K (p.Asn4Lys), gnomAD rs1972560240, REVEL 0.14, CADD 23.20
- V5L (p.Val5Leu), ExAC rs745363914, gnomAD rs745363914, REVEL 0.20, CADD 22.70
- D6G (p.Asp6Gly), Ensembl rs2123319592
- D6N (p.Asp6Asn), gnomAD rs1388963841, REVEL 0.48, CADD 25.40
- G7W (p.Gly7Trp), cosmic curated COSV99676, ExAC rs773936050
- L8P (p.Leu8Pro), TOPMed rs1428215749, gnomAD rs1428215749, REVEL 0.94, CADD 32.00
- Y11C (p.Tyr11Cys), rs748033766, ClinGen CA9513953, cosmic curated COSV55544, ClinVar RCV001136197, REVEL 0.58, CADD 25.20, Uncertain significance, Xeroderma pigmentosum, group D; not provided
- Y11F (p.Tyr11Phe), ExAC rs748033766, gnomAD rs748033766, REVEL 0.27, CADD 22.70, Uncertain significance
- Y11H (p.Tyr11His), ExAC rs777490688, TOPMed rs777490688, gnomAD rs777490688, REVEL 0.31, CADD 22.60
- P13Q (p.Pro13Gln), rs2514048618, ClinGen CA406380131, ClinVar RCV002366398, ClinVar RCV005931821, Uncertain significance, Inborn genetic diseases
- P13T (p.Pro13Thr), ExAC rs758518982, gnomAD rs758518982
- Y14* (p.Tyr14Ter), ESP rs141622611, TOPMed rs141622611, gnomAD rs141622611, CADD 37.00, Likely benign
- Y14C (p.Tyr14Cys), NCI-TCGA Cosmic COSV5554, cosmic curated COSV55540, Variant assessed as somatic; moderate impact.
- D15V (p.Asp15Val), rs2514048588, ClinGen CA406380093, ClinVar RCV004518415, Uncertain significance, Inborn genetic diseases
- Y16C (p.Tyr16Cys), rs147972150, ClinGen CA158761, ClinVar RCV000120770, ClinVar RCV000893772, REVEL 0.77, CADD 26.70, Conflicting interpretations, Ovarian cancer; not specified; not provided
- I17M (p.Ile17Met), rs1972558937, ClinGen CA406380046, ClinVar RCV004518418, Ensembl rs1972558937, AlphaMissense 0.42, MetaLR 0.83, Uncertain significance, Inborn genetic diseases
- P19A (p.Pro19Ala), rs1318658148, ClinGen CA406380027, ClinVar RCV002344880, REVEL 0.91, CADD 27.20, Uncertain significance, Inborn genetic diseases
- P19L (p.Pro19Leu), rs2514048540, ClinGen CA406380022, ClinVar RCV002347553, Uncertain significance, Inborn genetic diseases
- P19S (p.Pro19Ser), rs1318658148, ClinGen CA406380024, ClinVar RCV002344883, TOPMed rs1318658148, REVEL 0.90, CADD 28.90, Uncertain significance, Inborn genetic diseases
- E20A (p.Glu20Ala), ExAC rs761090656, gnomAD rs761090656, REVEL 0.75, CADD 31.00, Uncertain significance, Inborn genetic diseases
- E20K (p.Glu20Lys), rs764513844, ClinGen CA9513946, ClinVar RCV002355695, ClinVar RCV005626645, REVEL 0.80, CADD 31.00, Uncertain significance, Inborn genetic diseases; not provided
- Q21E (p.Gln21Glu), ExAC rs753306707, gnomAD rs753306707
- S23F (p.Ser23Phe), ExAC rs759037835, TOPMed rs759037835, gnomAD rs759037835, REVEL 0.62, CADD 26.00
- S23P (p.Ser23Pro), TOPMed rs1180365343, gnomAD rs1180365343, REVEL 0.46, CADD 24.40
- S23C (p.Ser23Cys), cosmic curated COSV55541, ExAC rs759037835, TOPMed rs759037835, gnomAD rs759037835
- S23T (p.Ser23Thr), TOPMed rs1180365343, gnomAD rs1180365343, REVEL 0.35, CADD 23.00
- S23del, rs886054500, Uncertain significance
- M25I (p.Met25Ile), Ensembl rs1972557729
- M25L (p.Met25Leu), rs773848568, ClinGen CA406379901, ClinVar RCV002380507, ClinGen CA9513941, AlphaMissense 0.48, MetaLR 0.88, Uncertain significance, Inborn genetic diseases
- M25R (p.Met25Arg), rs2123319234, ClinGen CA406379896, ClinVar RCV002046337, Ensembl rs2123319234, AlphaMissense 0.99, MetaLR 0.89, Uncertain significance, not provided
- M25V (p.Met25Val), ExAC rs773848568, TOPMed rs773848568, gnomAD rs773848568, Uncertain significance
- R26P (p.Arg26Pro), ExAC rs770507184, TOPMed rs770507184, gnomAD rs770507184, REVEL 0.35, CADD 23.20, Uncertain significance
- R26Q (p.Arg26Gln), rs770507184, ClinGen CA9513940, ClinVar RCV002409906, ExAC rs770507184, REVEL 0.15, CADD 22.60, Uncertain significance, Inborn genetic diseases
- R26W (p.Arg26Trp), rs933045867, ClinGen CA308975159, ClinVar RCV002400584, TOPMed rs933045867, REVEL 0.34, CADD 24.60, Uncertain significance, Inborn genetic diseases
- E27* (p.Glu27Ter), rs762622002, ClinGen CA9513939, ClinVar RCV003460028, ExAC rs762622002, CADD 38.00, Likely pathogenic
- E27G (p.Glu27Gly), Ensembl rs986893901
- L28R (p.Leu28Arg), Ensembl rs552042205
- K29E (p.Lys29Glu), rs1215067695, ClinGen CA406379877, ClinVar RCV001921040, ClinVar RCV002449585, REVEL 0.78, CADD 32.00, Uncertain significance, not provided; Inborn genetic diseases
- K29N (p.Lys29Asn), rs2514048407, ClinGen CA406379873, ClinVar RCV002373693, Uncertain significance, Inborn genetic diseases
- K29T (p.Lys29Thr), rs773018804, ClinGen CA9513938, ClinVar RCV002373411, ExAC rs773018804, REVEL 0.75, CADD 32.00, Uncertain significance, Inborn genetic diseases
- R30C (p.Arg30Cys), rs769614088, ClinGen CA9513937, ClinVar RCV003204417, ExAC rs769614088, REVEL 0.67, CADD 33.00, Uncertain significance, Inborn genetic diseases
- R30G (p.Arg30Gly), ExAC rs769614088, TOPMed rs769614088, gnomAD rs769614088, Uncertain significance
- T31M (p.Thr31Met), rs374798062, ClinGen CA9513936, ClinVar RCV002503254, ClinVar RCV003238717, REVEL 0.76, CADD 31.00, Uncertain significance, not provided; Cerebrooculofacioskeletal syndrome 2; Xeroderma pigmentosum, group
- T31R (p.Thr31Arg), ESP rs374798062, ExAC rs374798062, TOPMed rs374798062, gnomAD rs374798062, REVEL 0.81, CADD 31.00, Uncertain significance
- D33E (p.Asp33Glu), TOPMed rs1327800504, gnomAD rs1327800504, REVEL 0.61, CADD 24.30, Likely benign
- D33Y (p.Asp33Tyr), Ensembl rs1028669511
- A34P (p.Ala34Pro), rs768632615, ClinGen CA406379849, ClinVar RCV004525681, REVEL 0.48, CADD 32.00, Uncertain significance, Inborn genetic diseases
- A34T (p.Ala34Thr), rs768632615, ClinGen CA9513934, ClinVar RCV001927323, ClinVar RCV002490158, REVEL 0.27, CADD 25.40, Uncertain significance, Xeroderma pigmentosum, group D; Trichothiodystrophy 1, photosensitive; Cerebrooc
- A34V (p.Ala34Val), ExAC rs745939392, TOPMed rs745939392, gnomAD rs745939392, REVEL 0.29, CADD 23.90
- K35E (p.Lys35Glu), TOPMed rs1041573793, REVEL 0.24, CADD 24.40
- K35N (p.Lys35Asn), Ensembl rs1160897382
- K35R (p.Lys35Arg), Ensembl rs2123318952
- G36S (p.Gly36Ser), rs1972524741, ClinGen CA406379708, ClinVar RCV003278149, Ensembl rs1972524741, AlphaMissense 0.92, MetaLR 0.59, Uncertain significance, Inborn genetic diseases
- H37R (p.His37Arg), rs749368007, ClinGen CA9513909, ClinVar RCV001935016, ExAC rs749368007, REVEL 0.59, CADD 24.70, Uncertain significance, not provided
- G38R (p.Gly38Arg), Ensembl rs2123315103
- V39I (p.Val39Ile), rs778210446, ClinGen CA9513908, ClinVar RCV002373308, ExAC rs778210446, REVEL 0.14, CADD 19.50, Uncertain significance, Inborn genetic diseases
- L40P (p.Leu40Pro), rs1972524332, ClinGen CA406379646, ClinVar RCV002346921, Ensembl rs1972524332, REVEL 0.87, AlphaMissense 1.00, Uncertain significance, Inborn genetic diseases
- L40Q (p.Leu40Gln), rs1972524332, ClinGen CA406379648, ClinVar RCV004518340, AlphaMissense 1.00, MetaLR 0.81, Uncertain significance, Inborn genetic diseases
- E41* (p.Glu41Ter), rs1568546252, ClinGen CA406379637, ClinVar RCV000770818, Ensembl rs1568546252, Pathogenic
- E41G (p.Glu41Gly), rs2514045687, ClinGen CA406379634, ClinVar RCV004518343, Uncertain significance, Inborn genetic diseases
- P43L (p.Pro43Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S44L (p.Ser44Leu), NCI-TCGA Cosmic COSV5554, cosmic curated COSV55540, Ensembl rs2123315038, Variant assessed as somatic; moderate impact.
- T46I (p.Thr46Ile), NCI-TCGA Cosmic COSV5553, Variant assessed as somatic; moderate impact.
- T46N (p.Thr46Asn), rs2514045659, ClinGen CA2695198223, ClinVar RCV003467936, Likely pathogenic
- T46S (p.Thr46Ser), NCI-TCGA Cosmic COSV5553, cosmic curated COSV55538, Variant assessed as somatic; moderate impact.
- G47R (p.Gly47Arg), rs1360631927, ClinGen CA406379545, cosmic curated COSV55541, ClinVar RCV001531476, REVEL 0.96, CADD 27.70, Pathogenic, not provided; Cerebrooculofacioskeletal syndrome 2; Xeroderma pigmentosum, group
- V50I (p.Val50Ile), gnomAD rs1322143480, REVEL 0.24, CADD 19.70, Uncertain significance, Inborn genetic diseases
- L52P (p.Leu52Pro), rs752144394, ClinGen CA9513903, ClinVar RCV002405386, ExAC rs752144394, REVEL 0.82, CADD 29.00, Uncertain significance, Inborn genetic diseases
- L53W (p.Leu53Trp), rs2123314881, ClinGen CA406379491, cosmic curated COSV55545, ClinVar RCV001758571, AlphaMissense 0.98, MetaLR 0.84, Uncertain significance, not provided
- A54S (p.Ala54Ser), TOPMed rs992698178, gnomAD rs992698178, REVEL 0.30, AlphaMissense 0.43, Uncertain significance
- A54T (p.Ala54Thr), rs992698178, ClinGen CA406379484, cosmic curated COSV55540, ClinVar RCV002394820, AlphaMissense 0.43, MetaLR 0.24, Uncertain significance, Inborn genetic diseases
- L55P (p.Leu55Pro), rs587778274, ClinGen CA158800, ClinVar RCV000120783, ClinVar RCV002514632, REVEL 0.70, CADD 30.00, Uncertain significance, not provided
- L55V (p.Leu55Val), rs2514045576, ClinGen CA406379471, ClinVar RCV002403524, Uncertain significance, Inborn genetic diseases
- M57K (p.Met57Lys), ExAC rs746713272, gnomAD rs746713272, REVEL 0.48, CADD 24.40
- M57L (p.Met57Leu), rs2514045556, ClinGen CA406379445, ClinVar RCV002406281, Uncertain significance, Inborn genetic diseases
- Y59C (p.Tyr59Cys), rs1176128995, ClinGen CA406379409, ClinVar RCV001959698, TOPMed rs1176128995, REVEL 0.70, CADD 29.80, Uncertain significance, not provided
- Q60H (p.Gln60His), rs2514045522, ClinGen CA406379385, ClinVar RCV003278153, Uncertain significance, Inborn genetic diseases
- R61* (p.Arg61Ter), rs1420151470, ClinGen CA406379379, ClinVar RCV003550391, AlphaMissense 0.20, MetaLR 0.31, Pathogenic
- R61G (p.Arg61Gly), rs1420151470, ClinGen CA406379381, ClinVar RCV003733539, TOPMed rs1420151470, REVEL 0.31, AlphaMissense 0.20, Uncertain significance, not provided
- R61K (p.Arg61Lys), rs2514045505, ClinGen CA406379377, ClinVar RCV004518377, Uncertain significance, Inborn genetic diseases
- A62S (p.Ala62Ser), TOPMed rs1972518527
- A62V (p.Ala62Val), rs2514045108, ClinGen CA406379292, ClinVar RCV003147112, Uncertain significance, not provided
- Y63C (p.Tyr63Cys), rs373448214, ClinGen CA308974100, ClinVar RCV003204573, TOPMed rs373448214, REVEL 0.40, CADD 22.30, Uncertain significance, Inborn genetic diseases
- P64L (p.Pro64Leu), rs773453200, ClinGen CA9513872, cosmic curated COSV10583, ClinVar RCV002410669, REVEL 0.48, CADD 28.70, Uncertain significance, not provided; Inborn genetic diseases
- E66* (p.Glu66Ter), ExAC rs761965639, TOPMed rs761965639, gnomAD rs761965639, CADD 46.00, Pathogenic
- E66G (p.Glu66Gly), TOPMed rs961564676, gnomAD rs961564676, Uncertain significance
- E66V (p.Glu66Val), rs961564676, ClinGen CA308974085, ClinVar RCV002423647, ClinVar RCV005097866, REVEL 0.54, CADD 24.30, Uncertain significance, Inborn genetic diseases; not provided
- V67G (p.Val67Gly), Ensembl rs1599751089
- T68I (p.Thr68Ile), rs2514045007, ClinGen CA406379254, ClinVar RCV002419904, Uncertain significance, Inborn genetic diseases
- K69I (p.Lys69Ile), rs2514044992, ClinGen CA406379248, ClinVar RCV002297436, Uncertain significance, not provided
- L70H (p.Leu70His), Ensembl rs1357093006
- I71V (p.Ile71Val), NCI-TCGA Cosmic COSV9967, cosmic curated COSV99676, REVEL 0.14, CADD 21.00, Variant assessed as somatic; moderate impact.
- Y72C (p.Tyr72Cys), NCI-TCGA Cosmic COSV5553, cosmic curated COSV55538, NCI-TCGA Cosmic COSV9967, Variant assessed as somatic; moderate impact.
- Y72F (p.Tyr72Phe), NCI-TCGA Cosmic COSV5553, NCI-TCGA Cosmic COSV9967, cosmic curated COSV99676, Variant assessed as somatic; moderate impact.
- C73R (p.Cys73Arg), TOPMed rs1272175472
- C73Y (p.Cys73Tyr), TOPMed rs1972517345
- S74* (p.Ser74Ter), NCI-TCGA Cosmic COSV5553, NCI-TCGA Cosmic COSV5554, NCI-TCGA Cosmic COSV9967, cosmic curated COSV99676, Variant assessed as somatic; high impact.
- S74L (p.Ser74Leu), NCI-TCGA Cosmic COSV5553, cosmic curated COSV55538, NCI-TCGA Cosmic COSV5554, NCI-TCGA Cosmic COSV9967, Variant assessed as somatic; moderate impact.
- R75K (p.Arg75Lys), NCI-TCGA Cosmic COSV5554, cosmic curated COSV55544, Variant assessed as somatic; moderate impact.
- T76A (p.Thr76Ala), UniProt VAR 017282, Pathogenic, in XP-D
- V77L (p.Val77Leu), rs866646197, ClinGen CA406379154, ClinVar RCV002457541, TOPMed rs866646197, REVEL 0.32, CADD 22.70, Uncertain significance, Inborn genetic diseases
- V77M (p.Val77Met), rs866646197, ClinGen CA308974064, ClinVar RCV001136192, ClinVar RCV002429773, REVEL 0.24, CADD 23.00, Uncertain significance, Inborn genetic diseases; Xeroderma pigmentosum, group D
- P78S (p.Pro78Ser), rs373292179, ClinGen CA9513867, ClinVar RCV002448192, ClinVar RCV003098806, REVEL 0.42, CADD 23.00, Uncertain significance, Inborn genetic diseases; not provided
- I80T (p.Ile80Thr), NCI-TCGA Cosmic COSV5553, cosmic curated COSV55538, REVEL 0.69, CADD 23.80, Variant assessed as somatic; moderate impact.
- K82* (p.Lys82Ter), rs2514044862, ClinGen CA406379056, ClinVar RCV003572252, Pathogenic
- I84T (p.Ile84Thr), rs2514044139, ClinGen CA406378863, ClinVar RCV003172452, REVEL 0.65, CADD 24.00, Uncertain significance, Inborn genetic diseases
- I84V (p.Ile84Val), rs1254013195, ClinGen CA406378878, ClinVar RCV002024724, gnomAD rs1254013195, REVEL 0.18, CADD 20.30, Uncertain significance, not provided
- E85G (p.Glu85Gly), rs2514044117, ClinGen CA406378827, ClinVar RCV002928652, Uncertain significance, not provided
- E86* (p.Glu86Ter), rs2123313191, ClinVar RCV004576389, AlphaMissense 0.95, MetaLR 0.71, Likely pathogenic
- E86Q (p.Glu86Gln), NCI-TCGA Cosmic COSV5553, cosmic curated COSV55538, Ensembl rs2123313191, Variant assessed as somatic; moderate impact.
- L87I (p.Leu87Ile), rs2514044091, ClinGen CA406378788, ClinVar RCV002426199, cosmic curated COSV10806, Uncertain significance, Inborn genetic diseases
- L87P (p.Leu87Pro), rs779462120, ClinGen CA9513846, ClinVar RCV001528214, ClinVar RCV002424968, REVEL 0.84, CADD 30.00, Uncertain significance, Inborn genetic diseases; not provided
- R88* (p.Arg88Ter), rs748842373, ClinGen CA9513844, ClinVar RCV003236423, ClinVar RCV003466048, CADD 40.00, Pathogenic
- R88G (p.Arg88Gly), ExAC rs748842373, TOPMed rs748842373, gnomAD rs748842373, REVEL 0.55, CADD 23.50, Uncertain significance, not specified
- R88Q (p.Arg88Gln), rs777095373, ClinGen CA9513843, NCI-TCGA Cosmic COSV5554, cosmic curated COSV55544, REVEL 0.36, CADD 23.50, Uncertain significance, not provided
- K89E (p.Lys89Glu), rs2514044039, ClinGen CA406378754, ClinVar RCV003172454, REVEL 0.47, CADD 22.60, Uncertain significance, Inborn genetic diseases
- L90F (p.Leu90Phe), ExAC rs755818754, gnomAD rs755818754, REVEL 0.72, AlphaMissense 0.22
- L91H (p.Leu91His), rs1972509341, ClinGen CA406378685, ClinVar RCV004518405, AlphaMissense 0.87, MetaLR 0.55, Uncertain significance, Inborn genetic diseases
- L91P (p.Leu91Pro), cosmic curated COSV55539, Ensembl rs1972509341, REVEL 0.58, AlphaMissense 0.87
- N92K (p.Asn92Lys), rs982806873, ClinGen CA406378648, ClinVar RCV003172462, ClinGen CA406378651, REVEL 0.03, AlphaMissense 0.22, Uncertain significance, Inborn genetic diseases
- N92S (p.Asn92Ser), rs780965895, ClinGen CA9513840, ClinVar RCV000500978, ClinVar RCV002527246, REVEL 0.07, CADD 13.90, Conflicting interpretations, not specified; Inborn genetic diseases; not provided
- F93L (p.Phe93Leu), rs1328869143, ClinGen CA406378633, ClinVar RCV002441501, gnomAD rs1328869143, REVEL 0.45, CADD 22.60, Uncertain significance, Inborn genetic diseases
- Y94C (p.Tyr94Cys), ESP rs372410769, ExAC rs372410769, TOPMed rs372410769, gnomAD rs372410769, REVEL 0.49, CADD 23.20
- Y94H (p.Tyr94His), rs2514043964, ClinGen CA406378627, ClinVar RCV003358414, Uncertain significance, Inborn genetic diseases
- Y94S (p.Tyr94Ser), ESP rs372410769, ExAC rs372410769, TOPMed rs372410769, gnomAD rs372410769, REVEL 0.43, CADD 22.80
- E95D (p.Glu95Asp), TOPMed rs1281566631, gnomAD rs1281566631, REVEL 0.16, CADD 19.40
- E95G (p.Glu95Gly), rs571718677, ClinGen CA158803, cosmic curated COSV10583, ClinVar RCV000120784, REVEL 0.32, CADD 23.40, Benign/Likely benign, Xeroderma pigmentosum, group D; Cerebrooculofacioskeletal syndrome 2; Trichothio
- Q97L (p.Gln97Leu), rs762743220, ClinGen CA9513837, ClinVar RCV001933526, ClinVar RCV002441053, REVEL 0.25, CADD 23.00, Uncertain significance, Inborn genetic diseases; not provided
- E98D (p.Glu98Asp), rs145947678, ClinGen CA158806, ClinVar RCV000120785, ClinVar RCV000898560, REVEL 0.17, CADD 8.96, Benign/Likely benign, not provided; Xeroderma pigmentosum
- E98K (p.Glu98Lys), rs753975439, ClinGen CA9513836, cosmic curated COSV10941, ClinVar RCV002440047, REVEL 0.30, AlphaMissense 0.44, Uncertain significance, not provided; Inborn genetic diseases
- G99D (p.Gly99Asp), cosmic curated COSV10637, gnomAD rs1402868401, REVEL 0.58, CADD 23.00, Uncertain significance, Inborn genetic diseases
- E100* (p.Glu100Ter), rs964247601, ClinGen CA406378491, ClinVar RCV000770817, TOPMed rs964247601, AlphaMissense 0.06, MetaLR 0.36, Pathogenic
- E100K (p.Glu100Lys), rs964247601, ClinGen CA308973747, cosmic curated COSV55540, ClinVar RCV002442318, REVEL 0.37, AlphaMissense 0.06, Uncertain significance, Inborn genetic diseases
- K101N (p.Lys101Asn), rs1182986304, ClinGen CA406378446, ClinVar RCV002619801, ClinVar RCV003161958, REVEL 0.09, AlphaMissense 0.40, Uncertain significance, not provided; Inborn genetic diseases
- K101R (p.Lys101Arg), rs201123342, ClinGen CA406378459, ClinVar RCV002435975, 1000Genomes rs201123342, AlphaMissense 0.07, MetaLR 0.33, Uncertain significance, Inborn genetic diseases
- K101T (p.Lys101Thr), 1000Genomes rs201123342, ExAC rs201123342, gnomAD rs201123342, REVEL 0.28, AlphaMissense 0.07, Uncertain significance
- L102V (p.Leu102Val), Ensembl rs1018363931
- P103L (p.Pro103Leu), rs142462393, ClinGen CA9513832, cosmic curated COSV55540, ClinVar RCV000354908, REVEL 0.13, CADD 12.10, Uncertain significance, not provided; Xeroderma pigmentosum, group D
- P103Q (p.Pro103Gln), ESP rs142462393, ExAC rs142462393, TOPMed rs142462393, gnomAD rs142462393, REVEL 0.12, CADD 8.91, Uncertain significance
- P103R (p.Pro103Arg), rs142462393, ClinGen CA9513833, ClinVar RCV002770331, ESP rs142462393, REVEL 0.10, CADD 9.77, Uncertain significance, not provided
- G106E (p.Gly106Glu), rs2514043804, ClinGen CA406378243, ClinVar RCV004518407, REVEL 0.65, CADD 24.80, Uncertain significance, Inborn genetic diseases
- L107V (p.Leu107Val), gnomAD rs1212734412
- A108S (p.Ala108Ser), rs771447173, ClinGen CA406378202, ClinVar RCV002324733, REVEL 0.14, CADD 22.10, Uncertain significance, Inborn genetic diseases
- A108T (p.Ala108Thr), rs771447173, ClinGen CA9513830, ClinVar RCV002602683, ClinVar RCV003161882, REVEL 0.31, CADD 23.60, Uncertain significance, not provided; Inborn genetic diseases
- A108V (p.Ala108Val), rs1972507290, ClinGen CA406378189, ClinVar RCV004518408, TOPMed rs1972507290, REVEL 0.36, CADD 23.30, Uncertain significance, Inborn genetic diseases
- L109R (p.Leu109Arg), rs2514043674, ClinGen CA2695198222, ClinVar RCV003460024, REVEL 0.89, CADD 29.30, Uncertain significance, Inborn genetic diseases
- S110G (p.Ser110Gly), rs2514043745, ClinGen CA406378157, ClinVar RCV004518409, Uncertain significance, Inborn genetic diseases
- S110T (p.Ser110Thr), gnomAD rs1278299178, REVEL 0.26, CADD 20.90
- R112C (p.Arg112Cys), rs760820378, ClinGen CA9513829, cosmic curated COSV55539, ClinVar RCV001329857, REVEL 0.88, CADD 26.60, Conflicting interpretations, not specified; Trichothiodystrophy 1, photosensitive; Cerebrooculofacioskeletal
- R112G (p.Arg112Gly), 1000Genomes rs760820378, ExAC rs760820378, gnomAD rs760820378, REVEL 0.86, CADD 25.20, Uncertain significance, not specified
- R112H (p.Arg112His), rs121913020, ClinGen CA126883, cosmic curated COSV10454, ClinVar RCV000018273, REVEL 0.89, CADD 29.30, Pathogenic, not provided; Xeroderma pigmentosum, group D; Cerebrooculofacioskeletal syndrome
- K113N (p.Lys113Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- K113Q (p.Lys113Gln), rs2514043718, ClinGen CA406378102, ClinVar RCV003341839, Uncertain significance, Inborn genetic diseases
- N114H (p.Asn114His), Ensembl rs773632957, REVEL 0.62, CADD 26.60
- N114K (p.Asn114Lys), rs2514043687, ClinGen CA406378047, ClinVar RCV002337447, ClinGen CA406378036, Uncertain significance, Inborn genetic diseases
- L115F (p.Leu115Phe), rs2514043656, ClinGen CA406378013, ClinVar RCV002914390, Uncertain significance, not provided
- L115M (p.Leu115Met), rs2514043682, ClinGen CA406378033, ClinVar RCV002457116, Uncertain significance, Inborn genetic diseases
- L115S (p.Leu115Ser), Ensembl rs1435154200
- I117S (p.Ile117Ser), rs2514043641, ClinGen CA406377966, ClinVar RCV002459210, Uncertain significance, Inborn genetic diseases
- H118N (p.His118Asn), rs2514043633, ClinGen CA406377960, ClinVar RCV002459390, REVEL 0.30, CADD 22.90, Uncertain significance, Inborn genetic diseases
- H118Q (p.His118Gln), rs2514043619, ClinGen CA406377935, ClinVar RCV004518410, Uncertain significance, Inborn genetic diseases
- H118R (p.His118Arg), ExAC rs747684939, gnomAD rs747684939, REVEL 0.73, CADD 26.60
- H118Y (p.His118Tyr), rs2514043633, ClinGen CA406377953, ClinVar RCV002459393, NCI-TCGA Cosmic COSV5554, REVEL 0.63, CADD 28.60, Uncertain significance, Inborn genetic diseases
- P119A (p.Pro119Ala), rs2123312739, ClinGen CA406377933, ClinVar RCV001977797, Ensembl rs2123312739, REVEL 0.56, CADD 24.00, Uncertain significance, not provided
- E120D (p.Glu120Asp), gnomAD rs1349542172, REVEL 0.23, CADD 29.80
- E120Q (p.Glu120Gln), rs2514043593, ClinGen CA406377915, ClinVar RCV003839446, ClinVar RCV004621919, Uncertain significance, not provided; Inborn genetic diseases
- V121M (p.Val121Met), cosmic curated COSV55538, gnomAD rs1434217756, REVEL 0.77, CADD 32.00
- T122D (p.Thr122Asp), rs1235040517, ClinGen CA882711707, ClinVar RCV003727416, Pathogenic
- T122I (p.Thr122Ile), rs770334103, ClinGen CA9513811, ClinVar RCV002544201, ExAC rs770334103, REVEL 0.26, CADD 21.50, Uncertain significance, not provided
- P123A (p.Pro123Ala), rs994071519, ClinGen CA406376298, ClinVar RCV003306678, REVEL 0.34, AlphaMissense 0.06, Uncertain significance, Inborn genetic diseases
- P123L (p.Pro123Leu), rs747619345, ClinGen CA9513810, cosmic curated COSV10728, ClinVar RCV002346725, REVEL 0.28, CADD 22.30, Uncertain significance, Inborn genetic diseases
- P123T (p.Pro123Thr), rs994071519, ClinGen CA308970229, ClinVar RCV002452704, TOPMed rs994071519, AlphaMissense 0.06, MetaLR 0.10, Uncertain significance, Inborn genetic diseases
- L124V (p.Leu124Val), rs1406240724, ClinGen CA406376279, ClinVar RCV003165071, gnomAD rs1406240724, REVEL 0.41, CADD 15.60, Uncertain significance, Inborn genetic diseases
- R125C (p.Arg125Cys), rs372425466, ClinGen CA9513809, cosmic curated COSV10583, ClinVar RCV001900953, REVEL 0.78, CADD 32.00, Uncertain significance, not specified
- R125G (p.Arg125Gly), ESP rs372425466, ExAC rs372425466, TOPMed rs372425466, gnomAD rs372425466, REVEL 0.53, CADD 23.20, Uncertain significance
- R125H (p.Arg125His), rs746621981, ClinGen CA9513807, ClinVar RCV003088292, ClinVar RCV004073115, REVEL 0.60, CADD 23.20, Uncertain significance, Inborn genetic diseases; not provided
- G127R (p.Gly127Arg), rs2514035208, ClinGen CA406376224, ClinVar RCV003172431, Uncertain significance, Inborn genetic diseases
Public ERCC2 analysis runs
- ERCC2 analysis run — ERCC2 (1,693 variants) — completed 2026-08-18