CSF1R (P07333) variants and mutations
CSF1R (also known as P07333) is a human protein-coding gene encoding a macrophage colony-stimulating factor 1 receptor protein. Signals from CSF1 and IL-34 through this pathway are required for development, survival, and function of macrophages and microglia. Pathogenic variants can cause adult-onset leukoencephalopathy with cognitive, psychiatric, and motor deterioration. This analysis covers 2,023 CSF1R variants and mutations. Of these, 57% have computational variant effect predictions. Disease context includes leukoencephalopathy, diffuse hereditary, with spheroids 1, Hereditary diffuse leukoencephalopathy with axonal spheroids and pigmented glia, and brain abnormalities, neurodegeneration, and dysosteosclerosis. Example CSF1R variants include G2D, V5L, and L6P.
Variant analysis overview
- Gene: CSF1R
- Protein: P07333
- UniProt accession: P07333
- Organism: Homo sapiens
- Variants analyzed: 2023
- Variant scope: all variants
- Completed: 2026-08-18
Variant and mutation evidence
- Variant composition: 1,830 unspecified-consequence records; 1 stop retained variant; 8 frameshift variants; 54 missense variants; 12 in-frame deletions; 105 synonymous variants; 3 in-frame insertions; 5 splice-region variants; 2 stop-gained variants; 3 substitution
- Prediction scores: 1,143 variants have prediction scores (57% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: leukoencephalopathy, diffuse hereditary, with spheroids 1, Hereditary diffuse leukoencephalopathy with axonal spheroids and pigmented glia, brain abnormalities, neurodegeneration, and dysosteosclerosis, gastrointestinal stromal tumor, renal cell carcinoma, neoplasm, leukoencephalopathy, hereditary diffuse, with spheroids, tenosynovial giant cell tumor, diffuse type, neuroendocrine neoplasm, soft tissue sarcoma, sarcoma, tenosynovial giant cell tumor.
Protein structure and variant hotspots
- Protein features: 1 transmembrane segments; 6 domains; 2 binding sites; 20 post-translational modification sites.
- Structural context: 1,636 variants have structural context.
- PTM context: 44 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable CSF1R variants
Examples include G2D, V5L, L6P, L6V, L7M, L7R, L8F, V11M. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- G2D (p.Gly2Asp), cosmic curated COSV53840, TOPMed rs1758849369, CADD 15.30, PolyPhen-2 0.44
- V5L (p.Val5Leu), rs761624770, ClinGen CA3507322, ClinVar RCV000306661, ExAC rs761624770, CADD 6.18, PolyPhen-2 0.00, Likely benign, Hereditary diffuse leukoencephalopathy with spheroids
- L6P (p.Leu6Pro), gnomAD rs1423228852, CADD 17.20, PolyPhen-2 0.01
- L6V (p.Leu6Val), 1000Genomes rs544580321, gnomAD rs544580321, CADD 20.80, PolyPhen-2 0.15
- L7M (p.Leu7Met), gnomAD rs1351989543, CADD 22.30, PolyPhen-2 0.37
- L7R (p.Leu7Arg), 1000Genomes rs577425911, ExAC rs577425911, gnomAD rs577425911, CADD 26.40, PolyPhen-2 0.69
- L8F (p.Leu8Phe), Ensembl rs2113846037
- V11M (p.Val11Met), ExAC rs745892752, gnomAD rs745892752, CADD 15.30, PolyPhen-2 0.01
- A12G (p.Ala12Gly), gnomAD rs1183763649
- A12T (p.Ala12Thr), cosmic curated COSV53846, Ensembl rs2113846009
- A12V (p.Ala12Val), gnomAD rs1183763649, CADD 17.90, PolyPhen-2 0.00
- T13P (p.Thr13Pro), Ensembl rs2113845993
- A14D (p.Ala14Asp), NCI-TCGA Cosmic COSV5384, cosmic curated COSV53840, Variant assessed as somatic; moderate impact.
- A14G (p.Ala14Gly), ExAC rs774289908, gnomAD rs774289908, Uncertain significance
- A14V (p.Ala14Val), rs774289908, ClinGen CA3507318, ClinVar RCV003678296, ExAC rs774289908, CADD 13.60, PolyPhen-2 0.00, Uncertain significance, not provided
- W15C (p.Trp15Cys), Ensembl rs2113845969, CADD 29.10, PolyPhen-2 0.91
- W15R (p.Trp15Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H16L (p.His16Leu), Ensembl rs2113845955
- H16Y (p.His16Tyr), gnomAD rs1268162180
- G17A (p.Gly17Ala), Ensembl rs2113833772, CADD 17.30, PolyPhen-2 0.08
- Q18E (p.Gln18Glu), TOPMed rs1758518163, gnomAD rs1758518163, CADD 11.60, Uncertain significance, not provided
- G19A (p.Gly19Ala), cosmic curated COSV53843, Ensembl rs2113833763
- P21L (p.Pro21Leu), Ensembl rs2113833748, CADD 25.60, PolyPhen-2 1.00
- P21S (p.Pro21Ser), rs757795589, ClinGen CA3507291, cosmic curated COSV99036, ClinVar RCV001919088, CADD 25.90, PolyPhen-2 1.00, Uncertain significance, not provided
- P21T (p.Pro21Thr), ExAC rs757795589, TOPMed rs757795589, gnomAD rs757795589, CADD 25.50, PolyPhen-2 1.00, Uncertain significance
- I23T (p.Ile23Thr), ExAC rs749946644, gnomAD rs749946644, CADD 26.30, PolyPhen-2 1.00
- E24Q (p.Glu24Gln), rs1758517587, ClinGen CA361737936, ClinVar RCV003665458, Ensembl rs1758517587, CADD 16.90, PolyPhen-2 0.03, Uncertain significance, not provided
- S26N (p.Ser26Asn), gnomAD rs1188913271, CADD 9.14, PolyPhen-2 0.00
- V27I (p.Val27Ile), gnomAD rs1242725773
- V27L (p.Val27Leu), gnomAD rs1242725773
- P28S (p.Pro28Ser), NCI-TCGA TCGA novel, gnomAD rs1758517015, CADD 14.40, PolyPhen-2 0.07, Variant assessed as somatic; moderate impact.
- E29G (p.Glu29Gly), Ensembl rs1758516461
- E29K (p.Glu29Lys), ESP rs148727692, ExAC rs148727692, gnomAD rs148727692, CADD 22.50, PolyPhen-2 0.72
- E29Q (p.Glu29Gln), ESP rs148727692, ExAC rs148727692, gnomAD rs148727692, CADD 21.60
- L30Q (p.Leu30Gln), gnomAD rs1758516355, CADD 24.30, PolyPhen-2 1.00
- V31A (p.Val31Ala), NCI-TCGA Cosmic COSV5384, cosmic curated COSV53844, Variant assessed as somatic; moderate impact.
- V31D (p.Val31Asp), rs1758516240, ClinGen CA361737783, ClinVar RCV001767213, gnomAD rs1758516240, CADD 23.40, Uncertain significance, not provided
- V32A (p.Val32Ala), 1000Genomes rs56048668, ESP rs56048668, ExAC rs56048668, TOPMed rs56048668, CADD 23.70, PolyPhen-2 1.00, Benign
- V32G (p.Val32Gly), rs56048668, ClinGen CA3507281, cosmic curated COSV53839, ClinVar RCV000346339, CADD 24.00, PolyPhen-2 1.00, Benign/Likely benign, not specified; not provided; Hereditary diffuse leukoencephalopathy with spheroi
- V32L (p.Val32Leu), ESP rs372210450, ExAC rs372210450, TOPMed rs372210450, gnomAD rs372210450, Likely benign
- V32M (p.Val32Met), rs372210450, ClinGen CA3507282, cosmic curated COSV53832, ClinVar RCV002133914, CADD 23.20, PolyPhen-2 1.00, Conflicting interpretations, not provided; Inborn genetic diseases
- K33N (p.Lys33Asn), rs1229562677, gnomAD rs1229562677, NCI-TCGA Cosmic COSV5384, cosmic curated COSV53841, AlphaMissense 0.16, MetaLR 0.01, Variant assessed as somatic; moderate impact.
- P34A (p.Pro34Ala), Ensembl rs1758515301, CADD 15.40, PolyPhen-2 0.22
- P34L (p.Pro34Leu), TOPMed rs1381683092, gnomAD rs1381683092, CADD 22.90, PolyPhen-2 0.68
- P34S (p.Pro34Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G35A (p.Gly35Ala), gnomAD rs1397361181, CADD 22.50, PolyPhen-2 0.97, Uncertain significance
- G35E (p.Gly35Glu), rs1397361181, ClinGen CA361737717, ClinVar RCV002581646, gnomAD rs1397361181, CADD 22.80, PolyPhen-2 1.00, Uncertain significance, not provided
- G35R (p.Gly35Arg), TOPMed rs1331779557, gnomAD rs1331779557, CADD 23.10, PolyPhen-2 1.00
- A36S (p.Ala36Ser), Ensembl rs2113833625
- T37K (p.Thr37Lys), 1000Genomes rs139635308, ESP rs139635308, ExAC rs139635308, TOPMed rs139635308, CADD 0.47, PolyPhen-2 0.01, Uncertain significance
- T37M (p.Thr37Met), rs139635308, ClinGen CA3507280, cosmic curated COSV53828, ClinVar RCV002214913, CADD 1.31, PolyPhen-2 0.05, Conflicting interpretations, Brain abnormalities, neurodegeneration, and dysosteosclerosis; not provided
- V38E (p.Val38Glu), Ensembl rs2113833605
- T39A (p.Thr39Ala), Ensembl rs2113833598
- T39S (p.Thr39Ser), Ensembl rs2113833590
- R41* (p.Arg41Ter), cosmic curated COSV53828, TOPMed rs1391926262, gnomAD rs1391926262, CADD 35.00
- R41G (p.Arg41Gly), TOPMed rs1391926262, gnomAD rs1391926262, CADD 21.90, PolyPhen-2 0.95
- R41L (p.Arg41Leu), ExAC rs777239066, TOPMed rs777239066, gnomAD rs777239066, CADD 15.60, PolyPhen-2 0.16, Uncertain significance
- R41P (p.Arg41Pro), ExAC rs777239066, TOPMed rs777239066, gnomAD rs777239066, CADD 23.00, PolyPhen-2 0.98, Uncertain significance
- R41Q (p.Arg41Gln), rs777239066, ClinGen CA3507278, NCI-TCGA Cosmic COSV5384, cosmic curated COSV53842, CADD 21.20, PolyPhen-2 0.85, Uncertain significance, Inborn genetic diseases; not provided
- C42R (p.Cys42Arg), TOPMed rs1221129051, gnomAD rs1221129051, CADD 24.10, PolyPhen-2 1.00
- V43E (p.Val43Glu), Ensembl rs2113833563
- G44C (p.Gly44Cys), ESP rs147408195, ExAC rs147408195
- G44D (p.Gly44Asp), Ensembl rs2113833551
- G44S (p.Gly44Ser), ESP rs147408195, ExAC rs147408195
- N45I (p.Asn45Ile), Ensembl rs2113833538
- N45K (p.Asn45Lys), cosmic curated COSV53832, Ensembl rs2113833530
- G46A (p.Gly46Ala), Ensembl rs2113833524
- G46D (p.Gly46Asp), Ensembl rs2113833524
- S47G (p.Ser47Gly), ExAC rs774944970, gnomAD rs774944970, CADD 17.50, PolyPhen-2 0.18
- S47N (p.Ser47Asn), cosmic curated COSV10513, Ensembl rs2113833507, CADD 10.90, PolyPhen-2 0.01
- S47R (p.Ser47Arg), rs771756926, ExAC rs771756926, TOPMed rs771756926, gnomAD rs771756926, CADD 7.19, PolyPhen-2 0.80, Uncertain significance, Leukoencephalopathy, diffuse hereditary, with spheroids 1; not provided
- V48G (p.Val48Gly), Ensembl rs2113833483
- V48L (p.Val48Leu), TOPMed rs1256984931, gnomAD rs1256984931, CADD 18.90, PolyPhen-2 0.41, Likely benign
- V48M (p.Val48Met), rs1256984931, ClinGen CA361737165, NCI-TCGA Cosmic COSV5383, cosmic curated COSV53834, CADD 22.60, PolyPhen-2 0.69, Conflicting interpretations, not provided
- E49* (p.Glu49Ter), ExAC rs745585475, TOPMed rs745585475, gnomAD rs745585475, CADD 35.00, Uncertain significance
- E49D (p.Glu49Asp), ExAC rs778380548, gnomAD rs778380548, CADD 6.50, PolyPhen-2 0.00
- E49K (p.Glu49Lys), rs745585475, ClinGen CA3507273, NCI-TCGA Cosmic COSV5383, cosmic curated COSV53835, CADD 14.60, PolyPhen-2 0.00, Uncertain significance, Inborn genetic diseases
- W50C (p.Trp50Cys), ExAC rs756809440, gnomAD rs756809440
- W50G (p.Trp50Gly), Ensembl rs2113833466
- W50L (p.Trp50Leu), rs1561940695, ClinGen CA361737085, ClinVar RCV003556976, Ensembl rs1561940695, CADD 24.40, PolyPhen-2 1.00, Likely benign, not provided
- W50R (p.Trp50Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- D51E (p.Asp51Glu), TOPMed rs1206393347, gnomAD rs1206393347, CADD 0.04, PolyPhen-2 0.00
- G52A (p.Gly52Ala), ESP rs144261133, ExAC rs144261133, TOPMed rs144261133, gnomAD rs144261133
- G52D (p.Gly52Asp), NCI-TCGA Cosmic COSV9964, cosmic curated COSV99643, ESP rs144261133, ExAC rs144261133, Variant assessed as somatic; moderate impact.
- G52S (p.Gly52Ser), Ensembl rs2113833449
- G52V (p.Gly52Val), ESP rs144261133, ExAC rs144261133, TOPMed rs144261133, gnomAD rs144261133, CADD 14.20, PolyPhen-2 0.61
- P53A (p.Pro53Ala), TOPMed rs1433299442, gnomAD rs1433299442
- P53H (p.Pro53His), rs777789969, ClinGen CA361737001, ClinVar RCV001902413, ExAC rs777789969, AlphaMissense 0.07, MetaLR 0.01, Uncertain significance, not provided
- P53L (p.Pro53Leu), rs777789969, ClinGen CA3507269, NCI-TCGA Cosmic COSV9964, cosmic curated COSV99643, AlphaMissense 0.07, MetaLR 0.01, Uncertain significance, not provided
- P53S (p.Pro53Ser), TOPMed rs1433299442, gnomAD rs1433299442, CADD 8.72, PolyPhen-2 0.09
- P54H (p.Pro54His), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- P54Q (p.Pro54Gln), ExAC rs752543190, gnomAD rs752543190, CADD 3.82, PolyPhen-2 0.21
- P54R (p.Pro54Arg), ExAC rs752543190, gnomAD rs752543190, CADD 3.95, PolyPhen-2 0.12, Uncertain significance, Inborn genetic diseases
- P54S (p.Pro54Ser), ExAC rs755808680, TOPMed rs755808680, gnomAD rs755808680, CADD 0.03, PolyPhen-2 0.06, Likely benign, not provided
- P54T (p.Pro54Thr), ExAC rs755808680, TOPMed rs755808680, gnomAD rs755808680
- S55* (p.Ser55Ter), Ensembl rs2113833362
- P56A (p.Pro56Ala), Ensembl rs2113833357
- P56H (p.Pro56His), NCI-TCGA Cosmic COSV5382, NCI-TCGA Cosmic COSV5384, cosmic curated COSV53841, Variant assessed as somatic; moderate impact.
- P56L (p.Pro56Leu), Ensembl rs2113833352
- P56R (p.Pro56Arg), NCI-TCGA Cosmic COSV5382, cosmic curated COSV53828, NCI-TCGA Cosmic COSV5384, Variant assessed as somatic; moderate impact.
- P56S (p.Pro56Ser), cosmic curated COSV10458, NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H57Q (p.His57Gln), gnomAD rs1305733768, CADD 15.70, PolyPhen-2 0.32
- W58* (p.Trp58Ter), Ensembl rs2113833338, Pathogenic
- W58C (p.Trp58Cys), Ensembl rs2113833338
- W58R (p.Trp58Arg), ExAC rs767283490, TOPMed rs767283490, gnomAD rs767283490, CADD 23.30, PolyPhen-2 0.98, Uncertain significance, not provided
- T59I (p.Thr59Ile), Ensembl rs2113833328, CADD 10.40, PolyPhen-2 0.01
- T59S (p.Thr59Ser), Ensembl rs2113833334
- L60M (p.Leu60Met), 1000Genomes rs55865465, ExAC rs55865465, TOPMed rs55865465, gnomAD rs55865465, Benign
- L60P (p.Leu60Pro), rs1308547474, TOPMed rs1308547474, gnomAD rs1308547474, CADD 23.10, PolyPhen-2 0.97, Uncertain significance, not provided; Inborn genetic diseases
- L60V (p.Leu60Val), 1000Genomes rs55865465, ExAC rs55865465, TOPMed rs55865465, gnomAD rs55865465, CADD 7.71, PolyPhen-2 0.06, Benign
- Y61* (p.Tyr61Ter), NCI-TCGA Cosmic COSV5384, Variant assessed as somatic; high impact.
- Y61F (p.Tyr61Phe), Ensembl rs2113833300
- Y61H (p.Tyr61His), rs1423864756, NCI-TCGA Cosmic COSV5382, cosmic curated COSV53828, gnomAD rs1423864756, CADD 0.47, PolyPhen-2 0.01, Variant assessed as somatic; moderate impact.
- S62C (p.Ser62Cys), ExAC rs765380617, gnomAD rs765380617, CADD 13.60, PolyPhen-2 0.87
- D63G (p.Asp63Gly), Ensembl rs2113833283
- D63H (p.Asp63His), rs141621829, ClinGen CA3507258, ClinVar RCV001934043, ClinVar RCV003355678, CADD 19.70, PolyPhen-2 0.70, Conflicting interpretations, Inborn genetic diseases; not provided
- G64A (p.Gly64Ala), TOPMed rs1369244827, gnomAD rs1369244827, CADD 0.84
- G64D (p.Gly64Asp), TOPMed rs1369244827, gnomAD rs1369244827, CADD 4.32, PolyPhen-2 0.19
- G64V (p.Gly64Val), TOPMed rs1369244827, gnomAD rs1369244827, CADD 7.63, PolyPhen-2 0.19
- S65T (p.Ser65Thr), Ensembl rs2113833265
- S66G (p.Ser66Gly), rs760878957, ClinGen CA3507256, ClinVar RCV002030265, ExAC rs760878957, CADD 1.43, PolyPhen-2 0.01, Conflicting interpretations, not provided
- S66N (p.Ser66Asn), cosmic curated COSV53843, TOPMed rs1758508093, CADD 4.94, PolyPhen-2 0.08
- S66R (p.Ser66Arg), 1000Genomes rs536423346, ExAC rs536423346, TOPMed rs536423346, gnomAD rs536423346, CADD 3.01, PolyPhen-2 0.03
- S67N (p.Ser67Asn), rs147989288, ClinGen CA3507254, ClinVar RCV002003354, ClinVar RCV004752122, CADD 7.50, PolyPhen-2 0.05, Uncertain significance, not provided
- S67T (p.Ser67Thr), ESP rs147989288, ExAC rs147989288, TOPMed rs147989288, gnomAD rs147989288, Uncertain significance
- I68L (p.Ile68Leu), Ensembl rs2113833227
- I68S (p.Ile68Ser), gnomAD rs1288193831
- I68T (p.Ile68Thr), gnomAD rs1288193831, CADD 0.08, PolyPhen-2 0.01
- S70T (p.Ser70Thr), Ensembl rs2113833215
- T71N (p.Thr71Asn), gnomAD rs1259778590, CADD 21.10, PolyPhen-2 0.98
- T71S (p.Thr71Ser), gnomAD rs1259778590, CADD 20.60, PolyPhen-2 0.81
- N73D (p.Asn73Asp), gnomAD rs1351811725, CADD 20.60, PolyPhen-2 0.51
- A74P (p.Ala74Pro), ExAC rs756076440, TOPMed rs756076440, gnomAD rs756076440
- A74S (p.Ala74Ser), ExAC rs756076440, TOPMed rs756076440, gnomAD rs756076440, CADD 18.40, PolyPhen-2 0.59
- A74T (p.Ala74Thr), cosmic curated COSV53833, ExAC rs756076440, TOPMed rs756076440, gnomAD rs756076440, CADD 15.50, PolyPhen-2 0.20
- T75A (p.Thr75Ala), rs1325333723, ClinGen CA361736293, ClinVar RCV002893544, TOPMed rs1325333723, CADD 22.90, PolyPhen-2 0.77, Uncertain significance, Inborn genetic diseases
- T75I (p.Thr75Ile), rs748096324, ClinGen CA3507247, ClinVar RCV000351143, ClinVar RCV000890096, CADD 23.00, PolyPhen-2 0.99, Benign/Likely benign, Hereditary diffuse leukoencephalopathy with spheroids; not provided
- T75P (p.Thr75Pro), TOPMed rs1325333723, gnomAD rs1325333723, Uncertain significance
- T75S (p.Thr75Ser), TOPMed rs1325333723, gnomAD rs1325333723, CADD 14.70, PolyPhen-2 0.34, Uncertain significance
- F76L (p.Phe76Leu), Ensembl rs1758506093
- Q77E (p.Gln77Glu), TOPMed rs1487923086, Uncertain significance, Inborn genetic diseases
- N78T (p.Asn78Thr), Ensembl rs2113833125
- T79A (p.Thr79Ala), rs1014062385, NCI-TCGA Cosmic COSV9964, TOPMed rs1014062385, gnomAD rs1014062385, CADD 23.30, PolyPhen-2 0.93, Variant assessed as somatic; moderate impact.
- T79M (p.Thr79Met), rs1414323194, ClinGen CA361736159, cosmic curated COSV53834, ClinVar RCV003681464, CADD 22.60, PolyPhen-2 0.97, Uncertain significance, not provided
- T79P (p.Thr79Pro), NCI-TCGA Cosmic COSV9964, cosmic curated COSV99643, Variant assessed as somatic; moderate impact.
- T79R (p.Thr79Arg), gnomAD rs1414323194, CADD 23.70, PolyPhen-2 1.00, Uncertain significance
- T79S (p.Thr79Ser), TOPMed rs1014062385, gnomAD rs1014062385, CADD 23.00, PolyPhen-2 0.96
- G80W (p.Gly80Trp), rs2113833096, ClinGen CA361736143, ClinVar RCV002038874, Ensembl rs2113833096, CADD 18.70, PolyPhen-2 1.00, Uncertain significance, not provided
- T81S (p.Thr81Ser), Ensembl rs2113833086
- Y82C (p.Tyr82Cys), gnomAD rs1758505072, CADD 24.20
- Y82H (p.Tyr82His), Ensembl rs2113833075
- Y82S (p.Tyr82Ser), gnomAD rs1758505072
- R83C (p.Arg83Cys), cosmic curated COSV53838, ExAC rs753954924, TOPMed rs753954924, gnomAD rs753954924, CADD 23.70, PolyPhen-2 0.90
- R83G (p.Arg83Gly), ExAC rs753954924, TOPMed rs753954924, gnomAD rs753954924, CADD 22.80, PolyPhen-2 0.45
- R83H (p.Arg83His), rs761230419, ClinGen CA3507240, NCI-TCGA Cosmic COSV9964, cosmic curated COSV99643, CADD 0.71, PolyPhen-2 0.01, Uncertain significance, not provided
- R83L (p.Arg83Leu), ExAC rs761230419, TOPMed rs761230419, gnomAD rs761230419, CADD 7.23, PolyPhen-2 0.36, Uncertain significance
- R83S (p.Arg83Ser), ExAC rs753954924, TOPMed rs753954924, gnomAD rs753954924, CADD 16.30, PolyPhen-2 0.08
- C84S (p.Cys84Ser), Ensembl rs2113833043
- C84Y (p.Cys84Tyr), Ensembl rs2113833043
- T85I (p.Thr85Ile), rs1758504424, ClinVar RCV004576057, TOPMed rs1758504424, gnomAD rs1758504424, CADD 5.92, PolyPhen-2 0.56, Uncertain significance, not provided
- T85S (p.Thr85Ser), rs1402591976, ClinGen CA361736016, ClinVar RCV001952165, ClinVar RCV006352634, CADD 14.50, PolyPhen-2 0.17, Uncertain significance, Inborn genetic diseases; not provided
- E86D (p.Glu86Asp), rs767836397, ClinGen CA3507237, cosmic curated COSV10961, ClinVar RCV003353912, CADD 8.61, PolyPhen-2 0.44, Conflicting interpretations, Inborn genetic diseases; not provided
- E86G (p.Glu86Gly), Ensembl rs2113833022
- E86Q (p.Glu86Gln), ExAC rs775908212, TOPMed rs775908212, gnomAD rs775908212, CADD 18.80, PolyPhen-2 0.83, Uncertain significance, Inborn genetic diseases
- P87S (p.Pro87Ser), Ensembl rs2113833012
- G88* (p.Gly88Ter), Ensembl rs2113833007
- D89E (p.Asp89Glu), NCI-TCGA Cosmic COSV9964, cosmic curated COSV99643, ESP rs143080503, ExAC rs143080503, CADD 7.77, PolyPhen-2 0.00, Likely benign
- D89V (p.Asp89Val), Ensembl rs2113832996
- P90L (p.Pro90Leu), NCI-TCGA Cosmic COSV9964, cosmic curated COSV99641, Ensembl rs1758503493, CADD 17.40, PolyPhen-2 0.16, Variant assessed as somatic; moderate impact.
- P90T (p.Pro90Thr), rs150475750, ClinGen CA3507234, cosmic curated COSV99640, ClinVar RCV000371986, CADD 5.01, PolyPhen-2 0.01, Benign, not specified; not provided; Hereditary diffuse leukoencephalopathy with spheroi
- L91M (p.Leu91Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- L91R (p.Leu91Arg), rs762581670, ClinGen CA3507233, ClinVar RCV003024281, ExAC rs762581670, CADD 0.52, PolyPhen-2 0.00, Likely benign, not provided
- G92A (p.Gly92Ala), Ensembl rs2113832958, CADD 2.64, PolyPhen-2 0.00
- G93D (p.Gly93Asp), Ensembl rs2113832945
- G93S (p.Gly93Ser), ExAC rs772767792, CADD 3.95, PolyPhen-2 0.04
- A95T (p.Ala95Thr), cosmic curated COSV53830, TOPMed rs1437040009, gnomAD rs1437040009, CADD 15.30, PolyPhen-2 0.40, Likely benign, not provided
- A95V (p.Ala95Val), Ensembl rs2113832918
- A96T (p.Ala96Thr), rs1318254419, ClinGen CA361735696, NCI-TCGA Cosmic COSV5383, cosmic curated COSV53831, CADD 0.01, PolyPhen-2 0.00, Uncertain significance, not provided
- A96V (p.Ala96Val), NCI-TCGA Cosmic COSV9964, cosmic curated COSV99642, CADD 14.50, PolyPhen-2 0.00, Variant assessed as somatic; moderate impact.
- I97N (p.Ile97Asn), gnomAD rs1391078471
Public CSF1R analysis runs
- CSF1R analysis run — CSF1R (2,023 variants) — completed 2026-08-18