BMPR2 (Q13873) variants and mutations
BMPR2 (also known as Q13873) is a human protein-coding gene encoding a bone morphogenetic protein receptor type-2 protein. It initiates BMP signaling in vascular cells and helps maintain normal pulmonary-artery structure and endothelial function. Heterozygous loss-of-function variants are the most common known genetic cause of heritable pulmonary arterial hypertension. This analysis covers 1,426 BMPR2 variants and mutations. Of these, 69% have computational variant effect predictions. Disease context includes pulmonary hypertension, primary, 1, pulmonary arterial hypertension, and pulmonary venoocclusive disease. Example BMPR2 variants include T2S, T2A, and S3P.
Variant analysis overview
- Gene: BMPR2
- Protein: Q13873
- UniProt accession: Q13873
- Organism: Homo sapiens
- Variants analyzed: 1426
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 1,229 unspecified-consequence records; 94 missense variants; 79 synonymous variants; 7 splice-region variants; 3 in-frame deletions; 1 frameshift variants; 2 stop-gained variants; 10 substitution
- Prediction scores: 990 variants have prediction scores (69% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: pulmonary hypertension, primary, 1, pulmonary arterial hypertension, pulmonary venoocclusive disease, pulmonary venoocclusive disease 1, idiopathic pulmonary arterial hypertension, heritable pulmonary arterial hypertension, Pulmonary arterial hypertension associated with congenital heart disease, bone disorder, genetic non-acquired premature ovarian failure, spondylolisthesis, tibia fracture, spinal fusion.
Protein structure and variant hotspots
- Protein features: 1 transmembrane segments; 1 domains; 5 binding sites; 7 post-translational modification sites.
- Structural context: 412 variants have structural context.
- PTM context: 6 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable BMPR2 variants
Examples include T2S, T2A, S3P, S3S, S4L, S4S, L5P, L5R. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- T2S (p.Thr2Ser), TOPMed rs1690174370, REVEL 0.18, CADD 10.50, Uncertain significance, Pulmonary hypertension, primary, 1; Pulmonary venoocclusive disease 1
- T2A (p.Thr2Ala), gnomAD 2-202377478-A-G, REVEL 0.23, CADD 5.73
- S3P (p.Ser3Pro), ExAC rs748855275, gnomAD rs748855275, REVEL 0.27, CADD 13.90, Uncertain significance, Inborn genetic diseases
- S3S (p.Ser3Ser), rs549281044, gnomAD 2-202377483-C-A, CADD 9.89
- S4L (p.Ser4Leu), TOPMed rs922087863, gnomAD rs922087863, REVEL 0.34, CADD 23.00
- S4S (p.Ser4Ser), rs1255662189, gnomAD 2-202377486-G-A, CADD 13.90
- L5P (p.Leu5Pro), rs1690174755, ClinGen CA350396558, ClinVar RCV002389907, AlphaMissense 0.05, MetaLR 0.51, Uncertain significance, Inborn genetic diseases
- L5R (p.Leu5Arg), Ensembl rs1690174755, REVEL 0.35, AlphaMissense 0.05
- Q6* (p.Gln6Ter), rs886039219, ClinGen CA10587991, NCI-TCGA Cosmic COSV6581, cosmic curated COSV65812, Pathogenic
- Q6Q (p.Gln6Gln), gnomAD 2-202377492-G-A, CADD 12.30
- R7Q (p.Arg7Gln), TOPMed rs1167351312, gnomAD rs1167351312, REVEL 0.13, CADD 19.90
- R7G (p.Arg7Gly), gnomAD 2-202377493-C-G, REVEL 0.29, CADD 23.60
- R7R (p.Arg7Arg), rs774089439, gnomAD 2-202377493-C-A, CADD 14.10
- R7W (p.Arg7Trp), gnomAD 2-202377493-C-T, REVEL 0.37, CADD 24.20
- P8L (p.Pro8Leu), NCI-TCGA Cosmic COSV6581, cosmic curated COSV65813, REVEL 0.20, CADD 19.30, Variant assessed as somatic; moderate impact.
- P8T (p.Pro8Thr), gnomAD 2-202377496-C-A, REVEL 0.15, CADD 18.00
- P8S (p.Pro8Ser), gnomAD 2-202377496-C-T, REVEL 0.15, CADD 19.30
- W9* (p.Trp9Ter), rs1085307149, ClinGen CA350396608, NCI-TCGA Cosmic COSV6581, cosmic curated COSV65812, AlphaMissense 0.17, MetaLR 0.50, Pathogenic
- W9C (p.Trp9Cys), TOPMed rs1085307149, Pathogenic
- R10Q (p.Arg10Gln), rs761823322, ClinGen CA2060998, ClinVar RCV003596767, ClinVar RCV004369205, REVEL 0.12, CADD 22.10, Conflicting interpretations, Primary pulmonary hypertension; Inborn genetic diseases
- R10W (p.Arg10Trp), rs1085307150, ClinGen CA350396613, ClinVar RCV000488679, gnomAD rs1085307150, REVEL 0.17, CADD 23.70, Pathogenic, Pulmonary hypertension, primary, 1
- V11G (p.Val11Gly), Ensembl rs1574415812
- V11L (p.Val11Leu), ExAC rs767166903, TOPMed rs767166903, gnomAD rs767166903, REVEL 0.25, CADD 15.20
- V11V (p.Val11Val), rs906306607, gnomAD 2-202377507-G-A, CADD 13.60
- P12L (p.Pro12Leu), 1000Genomes rs373783006, ESP rs373783006, ExAC rs373783006, TOPMed rs373783006, REVEL 0.21, CADD 22.40
- P12P (p.Pro12Pro), gnomAD 2-202377510-C-T, CADD 13.90
- W13* (p.Trp13Ter), rs1085307152, ClinGen CA350396653, cosmic curated COSV10891, ClinVar RCV000488586, AlphaMissense 0.13, MetaLR 0.52, Pathogenic
- W13C (p.Trp13Cys), TOPMed rs1085307152, gnomAD rs1085307152, REVEL 0.23, AlphaMissense 0.13, Uncertain significance, Pulmonary hypertension, primary, 1; Pulmonary venoocclusive disease 1
- W13G (p.Trp13Gly), Ensembl rs1690175752
- W13S (p.Trp13Ser), gnomAD 2-202377512-G-C, REVEL 0.19, CADD 22.00
- L14V (p.Leu14Val), ExAC rs760946823, gnomAD rs760946823, REVEL 0.12, CADD 22.00
- L14L (p.Leu14Leu), gnomAD 2-202377516-A-C, CADD 10.20
- P15L (p.Pro15Leu), TOPMed rs1432200219, gnomAD rs1432200219, REVEL 0.17, CADD 15.90, Likely benign, Inborn genetic diseases
- P15P (p.Pro15Pro), rs1289095937, gnomAD 2-202377519-A-G, CADD 10.20
- W16* (p.Trp16Ter), rs1085307154, ClinGen CA350396691, NCI-TCGA Cosmic COSV6580, cosmic curated COSV65809, Pathogenic
- W16R (p.Trp16Arg), NCI-TCGA Cosmic COSV6580, cosmic curated COSV65809, Variant assessed as somatic; moderate impact.
- T17A (p.Thr17Ala), ExAC rs766753997, gnomAD rs766753997, REVEL 0.18, CADD 16.60
- T17S (p.Thr17Ser), ExAC rs766753997, gnomAD rs766753997, REVEL 0.15, CADD 16.10, Uncertain significance, Inborn genetic diseases
- T17N (p.Thr17Asn), gnomAD 2-202377524-C-A, REVEL 0.29, CADD 20.20
- I18M (p.Ile18Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- I18T (p.Ile18Thr), TOPMed rs1690176365
- I18V (p.Ile18Val), gnomAD 2-202377526-A-G, REVEL 0.17, CADD 11.90
- I18I (p.Ile18Ile), gnomAD 2-202377528-C-T, CADD 14.80
- L19L (p.Leu19Leu), gnomAD 2-202377529-C-T, CADD 14.80
- L20M (p.Leu20Met), TOPMed rs1365521743, gnomAD rs1365521743, REVEL 0.30, CADD 23.90
- L20L (p.Leu20Leu), rs765376013, gnomAD 2-202377534-G-A, CADD 14.40
- V21L (p.Val21Leu), gnomAD 2-202377535-G-C, REVEL 0.18, CADD 17.20
- V21V (p.Val21Val), rs149973695, gnomAD 2-202377537-C-T, CADD 15.00
- S22N (p.Ser22Asn), rs1227742705, gnomAD rs1227742705, REVEL 0.29, CADD 22.70, Variant assessed as somatic; moderate impact.
- S22G (p.Ser22Gly), gnomAD 2-202377538-A-G, REVEL 0.23, CADD 19.30
- S22T (p.Ser22Thr), gnomAD 2-202377539-G-C, REVEL 0.28, CADD 22.60
- S22S (p.Ser22Ser), rs1004254626, gnomAD 2-202377540-C-T, CADD 18.10
- T23A (p.Thr23Ala), rs141716313, ClinGen CA2061007, cosmic curated COSV10971, ClinVar RCV003596750, REVEL 0.34, CADD 7.67, Benign/Likely benign, Pulmonary hypertension, primary, 1; Pulmonary venoocclusive disease 1; Primary p
- T23I (p.Thr23Ile), rs140659948, ClinGen CA2061008, ClinVar RCV003082228, ClinVar RCV004963429, REVEL 0.21, CADD 19.50, Conflicting interpretations, Inborn genetic diseases; Primary pulmonary hypertension
- T23P (p.Thr23Pro), 1000Genomes rs141716313, ESP rs141716313, ExAC rs141716313, TOPMed rs141716313, Benign
- T23S (p.Thr23Ser), ESP rs140659948, ExAC rs140659948, TOPMed rs140659948, gnomAD rs140659948, REVEL 0.21, CADD 15.70, Uncertain significance, Inborn genetic diseases
- A24E (p.Ala24Glu), rs370120266, ClinGen CA2061011, NCI-TCGA Cosmic COSV6580, cosmic curated COSV65808, REVEL 0.39, CADD 22.90, Pathogenic, Pulmonary hypertension, primary, 1
- A24G (p.Ala24Gly), ESP rs370120266, ExAC rs370120266, TOPMed rs370120266, gnomAD rs370120266, REVEL 0.26, CADD 24.60, Pathogenic
- A24T (p.Ala24Thr), ESP rs377020025, ExAC rs377020025, TOPMed rs377020025, gnomAD rs377020025, REVEL 0.22, CADD 22.40, Uncertain significance, Inborn genetic diseases
- A24V (p.Ala24Val), ESP rs370120266, ExAC rs370120266, TOPMed rs370120266, gnomAD rs370120266, REVEL 0.23, CADD 21.50, Pathogenic
- A25V (p.Ala25Val), gnomAD 2-202377548-C-T, REVEL 0.20, CADD 23.20
- A25G (p.Ala25Gly), gnomAD 2-202377548-C-G, REVEL 0.20, CADD 23.20
- A25A (p.Ala25Ala), rs748943218, gnomAD 2-202377549-T-A, CADD 15.40
- A26E (p.Ala26Glu), rs1085307159, ClinGen CA350398932, ClinVar RCV000488646, Pathogenic
- A26A (p.Ala26Ala), gnomAD 2-202464810-T-C, CADD 15.50
- S27L (p.Ser27Leu), rs573463511, ClinGen CA2061031, cosmic curated COSV10100, ClinVar RCV003072388, REVEL 0.31, CADD 22.70, Conflicting interpretations, Inborn genetic diseases; Pulmonary hypertension, primary, 1; Pulmonary venoocclu
- S27S (p.Ser27Ser), rs147207234, gnomAD 2-202464813-G-A, CADD 4.88
- Q28* (p.Gln28Ter), rs1085307160, ClinGen CA350398957, ClinVar RCV000488714, Ensembl rs1085307160, Pathogenic
- Q28R (p.Gln28Arg), gnomAD 2-202464815-A-G, REVEL 0.56, CADD 23.50
- Q28Q (p.Gln28Gln), rs754688935, gnomAD 2-202464816-G-A, CADD 8.57
- N29S (p.Asn29Ser), rs112862820, ClinGen CA2061034, ClinVar RCV000389962, ClinVar RCV001507195, REVEL 0.28, CADD 16.80, Likely benign, Pulmonary arterial hypertension
- Q30* (p.Gln30Ter), rs1085307161, ClinGen CA350398991, ClinVar RCV000488840, ClinVar RCV006605272, Pathogenic
- Q30R (p.Gln30Arg), rs747740309, ClinGen CA2061035, ClinVar RCV003225679, ExAC rs747740309, AlphaMissense 0.08, MetaLR 0.81, Uncertain significance, Pulmonary hypertension, primary, 1
- Q30K (p.Gln30Lys), gnomAD 2-202464820-C-A, REVEL 0.33, CADD 23.00
- Q30P (p.Gln30Pro), gnomAD 2-202464821-A-C, REVEL 0.43, CADD 23.80
- Q30H (p.Gln30His), gnomAD 2-202464822-A-T, REVEL 0.40, CADD 23.10
- E31* (p.Glu31Ter), rs1085307162, ClinGen CA350399005, NCI-TCGA Cosmic COSV1010, ClinVar RCV000488591, AlphaMissense 0.22, MetaLR 0.86, Pathogenic
- E31G (p.Glu31Gly), Ensembl rs1692286705
- E31K (p.Glu31Lys), cosmic curated COSV10100, TOPMed rs1085307162, REVEL 0.50, AlphaMissense 0.22, Uncertain significance, not provided; Inborn genetic diseases
- R32Q (p.Arg32Gln), rs368430622, cosmic curated COSV10100, ESP rs368430622, ExAC rs368430622, REVEL 0.62, CADD 27.80, Uncertain significance, Pulmonary hypertension, primary, 1; Pulmonary venoocclusive disease 1; Inborn ge
- R32W (p.Arg32Trp), rs771887212, ExAC rs771887212, TOPMed rs771887212, gnomAD rs771887212, REVEL 0.72, CADD 30.00, Uncertain significance, Inborn genetic diseases
- L33L (p.Leu33Leu), rs1389564112, gnomAD 2-202464829-C-T, CADD 10.80
- L33I (p.Leu33Ile), gnomAD 2-202464829-C-A, REVEL 0.33, CADD 17.00
- C34R (p.Cys34Arg), rs1085307163, ClinGen CA350399040, ClinVar RCV000488668, ClinVar RCV001003649, AlphaMissense 1.00, MetaLR 0.99, Pathogenic, Pulmonary arterial hypertension
- A35R (p.Ala35Arg), rs1085307164, ClinGen CA645293989, ClinVar RCV000488842, Pathogenic
- A35T (p.Ala35Thr), TOPMed rs1692287185, Uncertain significance, Inborn genetic diseases
- A35V (p.Ala35Val), rs770128128, ClinGen CA64532180, NCI-TCGA Cosmic COSV6580, cosmic curated COSV65808, REVEL 0.57, CADD 25.90, Uncertain significance, Inborn genetic diseases; not provided
- A35A (p.Ala35Ala), rs746943205, gnomAD 2-202464837-G-A, CADD 10.80
- F36L (p.Phe36Leu), gnomAD 2-202464840-T-A, REVEL 0.71, CADD 23.10
- D38N (p.Asp38Asn), gnomAD 2-202464844-G-A, REVEL 0.58, CADD 27.60
- D38D (p.Asp38Asp), rs1304516739, gnomAD 2-202464846-T-C, CADD 10.30
- P39L (p.Pro39Leu), rs770804811, ClinGen CA2061039, cosmic curated COSV65809, ClinVar RCV003597107, REVEL 0.64, CADD 21.70, Conflicting interpretations, Primary pulmonary hypertension; Inborn genetic diseases
- P39R (p.Pro39Arg), rs1085307165, ClinGen CA645293990, ClinVar RCV000488570, Uncertain significance, Inborn genetic diseases
- P39S (p.Pro39Ser), cosmic curated COSV65808, TOPMed rs1341714453, gnomAD rs1341714453, REVEL 0.52, CADD 17.50
- P39P (p.Pro39Pro), rs776603012, gnomAD 2-202464849-G-A, CADD 2.13
- Y40* (p.Tyr40Ter), rs137852755, ClinGen CA119938, ClinVar RCV003984801, Ensembl rs137852755, Pathogenic
- Q41* (p.Gln41Ter), NCI-TCGA Cosmic COSV6580, cosmic curated COSV65809, Variant assessed as somatic; high impact.
- Q41H (p.Gln41His), Ensembl rs2105959678
- Q41R (p.Gln41Arg), gnomAD 2-202464854-A-G, REVEL 0.64, CADD 23.60
- Q41Q (p.Gln41Gln), gnomAD 2-202464855-G-A, CADD 5.28
- Q42* (p.Gln42Ter), rs1085307166, ClinGen CA350399161, ClinVar RCV000488756, Ensembl rs1085307166, Pathogenic
- Q42R (p.Gln42Arg), rs1085307167, ClinGen CA350399166, ClinVar RCV000488460, ClinVar RCV005051782, AlphaMissense 0.09, MetaLR 0.91, Uncertain significance, Pulmonary arterial hypertension
- Q42E (p.Gln42Glu), gnomAD 2-202464856-C-G, REVEL 0.54, CADD 17.70
- Q42Q (p.Gln42Gln), gnomAD 2-202464858-A-G, CADD 10.70
- D43A (p.Asp43Ala), gnomAD 2-202464860-A-C, REVEL 0.68, CADD 22.40
- L44L (p.Leu44Leu), gnomAD 2-202464864-T-C, CADD 12.40
- G45A (p.Gly45Ala), TOPMed rs1210216471, Uncertain significance, Inborn genetic diseases
- G45G (p.Gly45Gly), gnomAD 2-202464867-G-A, CADD 10.10
- I46L (p.Ile46Leu), cosmic curated COSV10748, ExAC rs759804753, TOPMed rs759804753, gnomAD rs759804753, REVEL 0.32, CADD 22.00, Likely benign, Primary pulmonary hypertension
- I46M (p.Ile46Met), TOPMed rs1692288256
- I46V (p.Ile46Val), rs759804753, ClinGen CA241419, ClinVar RCV000175688, ClinVar RCV002492748, REVEL 0.32, CADD 22.90, Uncertain significance, not provided; Pulmonary hypertension, primary, 1; Pulmonary venoocclusive diseas
- I46T (p.Ile46Thr), gnomAD 2-202464869-T-C, REVEL 0.51, CADD 21.10
- G47D (p.Gly47Asp), rs1085307168, ClinGen CA350399236, ClinVar RCV000488593, ClinVar RCV005051783, AlphaMissense 0.12, MetaLR 0.87, Uncertain significance, Pulmonary arterial hypertension
- G47S (p.Gly47Ser), TOPMed rs1692288347, REVEL 0.39, CADD 22.50
- E48D (p.Glu48Asp), NCI-TCGA TCGA novel, gnomAD rs1355532683, REVEL 0.56, CADD 19.80, Variant assessed as somatic; moderate impact.
- S49N (p.Ser49Asn), TOPMed rs1692288710, Uncertain significance, Inborn genetic diseases
- S49R (p.Ser49Arg), rs150080314, ClinGen CA2061042, ClinVar RCV002151984, ClinVar RCV004965779, REVEL 0.61, CADD 21.10, Conflicting interpretations, not provided; Primary pulmonary hypertension; Inborn genetic diseases
- S49S (p.Ser49Ser), rs150080314, gnomAD 2-202464879-T-C, CADD 13.90
- R50S (p.Arg50Ser), rs201759998, ClinGen CA350399269, ClinVar RCV003089746, ExAC rs201759998, REVEL 0.63, CADD 22.50, Likely benign, Primary pulmonary hypertension
- R50R (p.Arg50Arg), rs201759998, gnomAD 2-202464882-A-G, CADD 14.00
- I51L (p.Ile51Leu), TOPMed rs1466796813, gnomAD rs1466796813, REVEL 0.58, CADD 22.20, Uncertain significance, Inborn genetic diseases
- I51M (p.Ile51Met), TOPMed rs1692289098, gnomAD rs1692289098, REVEL 0.69, CADD 24.40, Uncertain significance, Inborn genetic diseases
- I51V (p.Ile51Val), TOPMed rs1466796813, gnomAD rs1466796813, REVEL 0.46, CADD 17.50, Uncertain significance, Inborn genetic diseases
- S52F (p.Ser52Phe), Ensembl rs1051805297, REVEL 0.53, CADD 20.90, Uncertain significance, Inborn genetic diseases
- S52S (p.Ser52Ser), gnomAD 2-202464888-T-G, CADD 13.20
- H53* (p.His53Ter), rs1085307169, ClinGen CA645293991, ClinVar RCV000488762, ClinVar RCV001003650, Pathogenic
- H53R (p.His53Arg), NCI-TCGA TCGA novel, REVEL 0.20, CADD 19.00, Uncertain significance, Inborn genetic diseases
- N55N (p.Asn55Asn), rs200976092, gnomAD 2-202464897-T-C, CADD 10.90
- G56A (p.Gly56Ala), TOPMed rs1282803122, Uncertain significance, Inborn genetic diseases
- G56R (p.Gly56Arg), gnomAD 2-202464898-G-A, REVEL 0.69, CADD 26.60
- G56G (p.Gly56Gly), rs1403322729, gnomAD 2-202464900-G-A, CADD 9.27
- T57Q (p.Thr57Gln), rs1085307170, ClinGen CA645293992, ClinVar RCV000488468, Pathogenic
- T57T (p.Thr57Thr), rs1395349205, gnomAD 2-202464903-A-T, CADD 10.30
- I58M (p.Ile58Met), ExAC rs752005716, gnomAD rs752005716, REVEL 0.43, CADD 23.00
- I58V (p.Ile58Val), TOPMed rs1692289613, Uncertain significance, Pulmonary hypertension, primary, 1; Pulmonary venoocclusive disease 1; Inborn ge
- L59del (p.Leu59del), gnomAD 2-202464904-ATAT-, CADD 19.30
- L59L (p.Leu59Leu), gnomAD 2-202464907-T-C, CADD 11.00
- C60F (p.Cys60Phe), rs1085307172, ClinGen CA350399336, ClinVar RCV001035315, Ensembl rs1085307172, AlphaMissense 0.99, MetaLR 0.98, Uncertain significance, Pulmonary hypertension, primary, 1
- C60G (p.Cys60Gly), rs1085307171, ClinGen CA350399333, ClinVar RCV000488815, Ensembl rs1085307171, AlphaMissense 1.00, MetaLR 0.97, Pathogenic, Pulmonary hypertension, primary, 1
- C60R (p.Cys60Arg), rs1085307171, ClinGen CA350399332, ClinVar RCV000488650, Ensembl rs1085307171, AlphaMissense 1.00, MetaLR 0.97, Pathogenic, Pulmonary hypertension, primary, 1
- C60Y (p.Cys60Tyr), rs1085307172, ClinGen CA350399334, ClinVar RCV000488506, UniProt VAR 013670, AlphaMissense 0.99, MetaLR 0.98, Pathogenic, Pulmonary hypertension, primary, 1
- C60C (p.Cys60Cys), rs2105959771, gnomAD 2-202464912-C-T, CADD 8.66
- S61L (p.Ser61Leu), rs1166280962, ClinGen CA350399344, ClinVar RCV003050521, ClinVar RCV005028142, REVEL 0.43, CADD 22.00, Conflicting interpretations, Inborn genetic diseases; Primary pulmonary hypertension; Pulmonary hypertension
- S61P (p.Ser61Pro), gnomAD rs1692289934, REVEL 0.56, CADD 22.20
- S61T (p.Ser61Thr), NCI-TCGA Cosmic COSV6581, cosmic curated COSV65810, Variant assessed as somatic; moderate impact.
- S61W (p.Ser61Trp), gnomAD 2-202464914-C-G, REVEL 0.66, CADD 25.20
- S61S (p.Ser61Ser), rs762330274, gnomAD 2-202464915-G-A, CADD 9.06
- K62E (p.Lys62Glu), TOPMed rs1324547976, gnomAD rs1324547976, REVEL 0.52, CADD 22.40, Uncertain significance, Inborn genetic diseases
- K62T (p.Lys62Thr), gnomAD 2-202464917-A-C, REVEL 0.76, CADD 24.10
- G63R (p.Gly63Arg), rs767827692, ClinGen CA2061048, ClinVar RCV003283199, ExAC rs767827692, REVEL 0.86, CADD 27.10, Uncertain significance, Inborn genetic diseases
- G63Y (p.Gly63Tyr), rs1553503200, ClinGen CA645293993, ClinVar RCV000488633, Pathogenic
- G63fsX1, rs863223423, Pathogenic
- S64* (p.Ser64Ter), rs2469639019, ClinGen CA2580065450, ClinVar RCV002285241, ClinVar RCV006470429, Pathogenic, in PPH1
- S64G (p.Ser64Gly), TOPMed rs1391212374, REVEL 0.59, CADD 22.50, Uncertain significance, in PPH1
- S64I (p.Ser64Ile), Ensembl rs1692290460, REVEL 0.71, CADD 25.60, Uncertain significance, Inborn genetic diseases
- S64R (p.Ser64Arg), UniProt VAR 079588, Uncertain significance, in PPH1
- S64N (p.Ser64Asn), gnomAD 2-202464923-G-A, REVEL 0.44, CADD 22.70
- S64S (p.Ser64Ser), rs750825305, gnomAD 2-202464924-C-T, CADD 12.40
- T65S (p.Thr65Ser), gnomAD rs1348032578
- T65I (p.Thr65Ile), gnomAD 2-202464926-C-T, REVEL 0.35, CADD 17.10
- C66G (p.Cys66Gly), rs1085307175, ClinGen CA350399374, ClinVar RCV000488793, Ensembl rs1085307175, AlphaMissense 1.00, MetaLR 1.00, Pathogenic, Pulmonary hypertension, primary, 1
- C66R (p.Cys66Arg), rs1085307175, ClinGen CA350399373, ClinVar RCV000488696, Ensembl rs1085307175, AlphaMissense 1.00, MetaLR 1.00, Pathogenic, Pulmonary hypertension, primary, 1
- C66Y (p.Cys66Tyr), rs1085307176, ClinGen CA350399375, ClinVar RCV000488535, Ensembl rs1085307176, AlphaMissense 1.00, MetaLR 1.00, Pathogenic, Pulmonary hypertension, primary, 1
- Y67* (p.Tyr67Ter), rs1085307179, ClinGen CA350399387, ClinVar RCV000488520, ClinVar RCV001376584, Pathogenic, in PPH1
- Y67C (p.Tyr67Cys), rs1085307177, ClinGen CA350399384, cosmic curated COSV10100, ClinVar RCV000488664, REVEL 0.89, CADD 24.80, Pathogenic, Primary pulmonary hypertension; Pulmonary hypertension, primary, 1
- Y67H (p.Tyr67His), rs1559046623, ClinGen CA350399381, cosmic curated COSV65812, ClinVar RCV000755850, AlphaMissense 0.94, MetaLR 0.93, Uncertain significance, not provided
- G68D (p.Gly68Asp), rs1085307180, ClinGen CA350399390, cosmic curated COSV65809, ClinVar RCV000488700, AlphaMissense 1.00, MetaLR 0.96, Pathogenic, Pulmonary hypertension, primary, 1; Pulmonary arterial hypertension
- G68S (p.Gly68Ser), ExAC rs754561255, gnomAD rs754561255
- W70* (p.Trp70Ter), NCI-TCGA Cosmic COSV1010, cosmic curated COSV10100, Variant assessed as somatic; high impact.
- E71A (p.Glu71Ala), ExAC rs778682407, TOPMed rs778682407, gnomAD rs778682407, REVEL 0.86, CADD 24.20
- E71K (p.Glu71Lys), rs1553503208, ClinGen CA350399408, cosmic curated COSV10468, ClinVar RCV000664171, REVEL 0.75, CADD 23.00, Uncertain significance, Pulmonary arterial hypertension associated with congenital heart disease
- E71Q (p.Glu71Gln), gnomAD 2-202464943-G-C, REVEL 0.72, CADD 23.90
- K72R (p.Lys72Arg), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S73* (p.Ser73Ter), rs137852742, ClinGen CA278072, ClinVar RCV000009342, ClinVar RCV001003653, AlphaMissense 0.13, MetaLR 0.87, Pathogenic
- S73L (p.Ser73Leu), gnomAD rs137852742, REVEL 0.36, AlphaMissense 0.13, Pathogenic
- S73T (p.Ser73Thr), TOPMed rs1364793883, gnomAD rs1364793883, REVEL 0.33, CADD 17.60
- S73S (p.Ser73Ser), rs752139986, gnomAD 2-202464951-A-G, CADD 9.43
- K74E (p.Lys74Glu), rs757855256, ClinGen CA2061053, ClinVar RCV000983865, ClinVar RCV002427435, REVEL 0.35, CADD 19.60, Likely benign, Pulmonary arterial hypertension
- G75A (p.Gly75Ala), ExAC rs777451350, TOPMed rs777451350, gnomAD rs777451350, REVEL 0.92, CADD 25.60, Uncertain significance, Inborn genetic diseases
- G75E (p.Gly75Glu), NCI-TCGA Cosmic COSV6580, cosmic curated COSV65807, REVEL 0.91, CADD 26.20, Variant assessed as somatic; moderate impact.
Public BMPR2 analysis runs
- BMPR2 analysis run — BMPR2 (1,426 variants) — completed 2026-08-21