ATXN1 (Ataxin-1) variants and mutations
ATXN1 (also known as Ataxin-1) is a human protein-coding gene encoding an ataxin-1 protein. It participates in nuclear transcriptional and RNA-regulatory complexes in neurons. Expansion of its polyglutamine tract causes spinocerebellar ataxia type 1 through a toxic gain of function that progressively injures cerebellar and brainstem neurons. This analysis covers 1,547 ATXN1 variants and mutations. Of these, 76% have computational variant effect predictions. Disease context includes spinocerebellar ataxia type 1, schizophrenia, and intelligence. Example ATXN1 variants include K2R, N4I, and N4S.
Variant analysis overview
- Gene: ATXN1
- Protein: Ataxin-1
- UniProt accession: P54253
- Organism: Homo sapiens
- Variants analyzed: 1547
- Variant scope: all variants
- Completed: 2026-08-22
Variant and mutation evidence
- Variant composition: 1,100 unspecified-consequence records; 218 synonymous variants; 214 missense variants; 11 frameshift variants; 1 in-frame deletions; 2 stop-gained variants; 1 splice-region variants
- Prediction scores: 1,174 variants have prediction scores (76% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: spinocerebellar ataxia type 1, schizophrenia, intelligence, atrial fibrillation, systemic lupus erythematosus, androgenetic alopecia, plasma cell myeloma, intestinal disorder, stomach disorder, vitiligo, multiple sclerosis, Back pain.
Protein structure and variant hotspots
- Protein features: 1 domains; 5 post-translational modification sites.
- Structural context: 266 variants have structural context.
- PTM context: 11 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable ATXN1 variants
Examples include K2R, N4I, N4S, N4Y, Q5*, E6Q, R7L, R7W. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- K2R (p.Lys2Arg), ExAC rs758505326, TOPMed rs758505326, gnomAD rs758505326
- N4I (p.Asn4Ile), ExAC rs748241978, TOPMed rs748241978, gnomAD rs748241978, REVEL 0.17, CADD 22.80
- N4S (p.Asn4Ser), ExAC rs748241978, TOPMed rs748241978, gnomAD rs748241978, REVEL 0.16, CADD 17.60
- N4Y (p.Asn4Tyr), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99784, Variant assessed as somatic; moderate impact.
- Q5* (p.Gln5Ter), NCI-TCGA Cosmic COSV5521, cosmic curated COSV55219, AlphaMissense 0.54, CADD 12.30, Variant assessed as somatic; high impact.
- E6Q (p.Glu6Gln), NCI-TCGA Cosmic COSV5521, cosmic curated COSV55213, Variant assessed as somatic; moderate impact.
- R7L (p.Arg7Leu), NCI-TCGA TCGA novel, TOPMed rs1760897417, Variant assessed as somatic; moderate impact.
- R7W (p.Arg7Trp), NCI-TCGA TCGA novel, TOPMed rs1760897481, gnomAD rs1760897481, REVEL 0.39, CADD 26.30, Variant assessed as somatic; moderate impact.
- S8N (p.Ser8Asn), cosmic curated COSV55208, gnomAD rs1316779489, REVEL 0.23, CADD 23.60
- N9K (p.Asn9Lys), ExAC rs759716662, TOPMed rs759716662, gnomAD rs759716662, REVEL 0.15, AlphaMissense 0.20
- E10K (p.Glu10Lys), cosmic curated COSV55231, REVEL 0.32, CADD 24.60
- C11R (p.Cys11Arg), ExAC rs753921403, gnomAD rs753921403
- C11S (p.Cys11Ser), TOPMed rs1245185054
- C11Y (p.Cys11Tyr), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99787, Variant assessed as somatic; moderate impact.
- P13S (p.Pro13Ser), NCI-TCGA Cosmic COSV5520, cosmic curated COSV55208, REVEL 0.48, AlphaMissense 0.39, Variant assessed as somatic; moderate impact.
- R17C (p.Arg17Cys), NCI-TCGA TCGA novel, REVEL 0.38, CADD 27.70, Variant assessed as somatic; moderate impact.
- R17H (p.Arg17His), TOPMed rs1250580364, REVEL 0.37, AlphaMissense 0.18
- E18G (p.Glu18Gly), cosmic curated COSV10504, REVEL 0.29, CADD 28.10
- I19T (p.Ile19Thr), Ensembl rs75068405, REVEL 0.38, AlphaMissense 0.14
- P20L (p.Pro20Leu), gnomAD rs1366944802, REVEL 0.13, AlphaMissense 0.15
- A21P (p.Ala21Pro), ExAC rs774113311, TOPMed rs774113311, gnomAD rs774113311, REVEL 0.24, AlphaMissense 0.32
- A21T (p.Ala21Thr), cosmic curated COSV55212, ExAC rs774113311, TOPMed rs774113311, gnomAD rs774113311, REVEL 0.21, AlphaMissense 0.32
- T22P (p.Thr22Pro), ExAC rs748739614, gnomAD rs748739614, REVEL 0.15, CADD 23.60
- S23R (p.Ser23Arg), TOPMed rs1301516493, gnomAD rs1301516493, REVEL 0.17, AlphaMissense 0.33
- R24P (p.Arg24Pro), cosmic curated COSV55221, REVEL 0.10, CADD 23.80
- R24Q (p.Arg24Gln), TOPMed rs1189003389, gnomAD rs1189003389, REVEL 0.10, CADD 23.20
- R24W (p.Arg24Trp), rs1394208682, gnomAD rs1394208682, REVEL 0.13, CADD 26.80, Variant assessed as somatic; moderate impact.
- S25Y (p.Ser25Tyr), TOPMed rs1424936726, REVEL 0.15, CADD 23.40
- S26C (p.Ser26Cys), cosmic curated COSV55207
- S26F (p.Ser26Phe), cosmic curated COSV55208
- E27G (p.Glu27Gly), 1000Genomes rs139225641, ExAC rs139225641, gnomAD rs139225641, REVEL 0.10, CADD 26.40
- E27K (p.Glu27Lys), cosmic curated COSV99784, 1000Genomes rs551689167, TOPMed rs551689167, gnomAD rs551689167, REVEL 0.12, AlphaMissense 0.07
- E27Q (p.Glu27Gln), 1000Genomes rs551689167, TOPMed rs551689167, gnomAD rs551689167, REVEL 0.15, AlphaMissense 0.10
- E27V (p.Glu27Val), cosmic curated COSV10584
- E28D (p.Glu28Asp), TOPMed rs1760895460, gnomAD rs1760895460, REVEL 0.07, AlphaMissense 0.43
- A30S (p.Ala30Ser), cosmic curated COSV55211, TOPMed rs1760895329, REVEL 0.04, AlphaMissense 0.07
- P31A (p.Pro31Ala), gnomAD rs1212904671, REVEL 0.03, CADD 0.74
- T32I (p.Thr32Ile), 1000Genomes rs150375774, ESP rs150375774, ExAC rs150375774, TOPMed rs150375774, REVEL 0.06, AlphaMissense 0.09, Benign
- T32N (p.Thr32Asn), 1000Genomes rs150375774, ESP rs150375774, ExAC rs150375774, TOPMed rs150375774, Benign
- T32P (p.Thr32Pro), Ensembl rs1581693065
- T32S (p.Thr32Ser), rs150375774, ClinGen CA3645719, ClinVar RCV001356166, 1000Genomes rs150375774, AlphaMissense 0.09, MetaLR 0.02, Benign, not provided
- S35N (p.Ser35Asn), gnomAD rs1229618656, REVEL 0.08, AlphaMissense 0.21
- S35R (p.Ser35Arg), ESP rs140257227, ExAC rs140257227, TOPMed rs140257227, gnomAD rs140257227, REVEL 0.04, CADD 19.80
- N37S (p.Asn37Ser), ExAC rs766480685, TOPMed rs766480685, gnomAD rs766480685, REVEL 0.10, CADD 15.90
- H38Q (p.His38Gln), Ensembl rs2113415069, REVEL 0.10, CADD 18.70
- R39L (p.Arg39Leu), cosmic curated COSV55226, ExAC rs764254890, TOPMed rs764254890, gnomAD rs764254890, REVEL 0.13, CADD 23.20
- R39P (p.Arg39Pro), ExAC rs764254890, TOPMed rs764254890, gnomAD rs764254890, REVEL 0.16, CADD 25.00
- R39Q (p.Arg39Gln), rs764254890, NCI-TCGA Cosmic COSV5522, cosmic curated COSV55221, REVEL 0.07, CADD 23.50, Uncertain significance, Inborn genetic diseases
- R39W (p.Arg39Trp), rs1379316974, NCI-TCGA Cosmic COSV5522, cosmic curated COSV55221, gnomAD rs1379316974, REVEL 0.18, CADD 24.50, Variant assessed as somatic; moderate impact.
- V40A (p.Val40Ala), gnomAD rs1168923062, REVEL 0.03, CADD 14.30
- V40M (p.Val40Met), ExAC rs761735732, gnomAD rs761735732, REVEL 0.05, CADD 22.30
- E41D (p.Glu41Asp), cosmic curated COSV99068
- G42A (p.Gly42Ala), ESP rs146653003, ExAC rs146653003, TOPMed rs146653003, gnomAD rs146653003, REVEL 0.02, CADD 19.00, Likely benign, not provided
- G42D (p.Gly42Asp), cosmic curated COSV55221, ESP rs146653003, ExAC rs146653003, TOPMed rs146653003, REVEL 0.02, CADD 16.10
- T43I (p.Thr43Ile), gnomAD rs1168661269
- A44P (p.Ala44Pro), gnomAD rs1760893886, REVEL 0.09, AlphaMissense 0.30
- A44T (p.Ala44Thr), NCI-TCGA TCGA novel, REVEL 0.03, AlphaMissense 0.08, Uncertain significance, Inborn genetic diseases
- A44V (p.Ala44Val), cosmic curated COSV55220, Ensembl rs1581692998, REVEL 0.11, AlphaMissense 0.17
- W45* (p.Trp45Ter), gnomAD rs1414571635, CADD 36.00
- W45R (p.Trp45Arg), TOPMed rs1760893763
- P47L (p.Pro47Leu), cosmic curated COSV55211, ExAC rs775100540, TOPMed rs775100540, gnomAD rs775100540, REVEL 0.12, AlphaMissense 0.45, Uncertain significance, Inborn genetic diseases
- P47S (p.Pro47Ser), cosmic curated COSV55208, REVEL 0.14, AlphaMissense 0.45
- G48C (p.Gly48Cys), gnomAD rs1206306975
- G48D (p.Gly48Asp), gnomAD rs1484269896, REVEL 0.10, CADD 17.50
- N49K (p.Asn49Lys), ExAC rs778398422, TOPMed rs778398422, gnomAD rs778398422, REVEL 0.07, AlphaMissense 0.36
- P50T (p.Pro50Thr), ExAC rs772316456, gnomAD rs772316456
- G52V (p.Gly52Val), gnomAD rs1321973842, REVEL 0.03, CADD 16.80, Uncertain significance, Inborn genetic diseases
- R53G (p.Arg53Gly), ExAC rs779170808, TOPMed rs779170808, gnomAD rs779170808, REVEL 0.06, CADD 23.70
- R53L (p.Arg53Leu), ExAC rs754100060, TOPMed rs754100060, gnomAD rs754100060, REVEL 0.01, CADD 16.60, Uncertain significance, Inborn genetic diseases
- R53P (p.Arg53Pro), ExAC rs754100060, TOPMed rs754100060, gnomAD rs754100060, REVEL 0.04, CADD 20.70, Likely benign
- R53Q (p.Arg53Gln), ExAC rs754100060, TOPMed rs754100060, gnomAD rs754100060, REVEL 0.03, CADD 15.00, Uncertain significance, Inborn genetic diseases
- R53W (p.Arg53Trp), cosmic curated COSV10960, ExAC rs779170808, TOPMed rs779170808, gnomAD rs779170808, REVEL 0.12, CADD 24.90, Uncertain significance, Inborn genetic diseases
- G54A (p.Gly54Ala), ExAC rs762985181, TOPMed rs762985181, gnomAD rs762985181
- G54D (p.Gly54Asp), ExAC rs762985181, TOPMed rs762985181, gnomAD rs762985181, REVEL 0.11, AlphaMissense 0.52
- H55L (p.His55Leu), ExAC rs756245803, TOPMed rs756245803, gnomAD rs756245803, REVEL 0.03, CADD 11.70
- H55P (p.His55Pro), ExAC rs756245803, TOPMed rs756245803, gnomAD rs756245803, REVEL 0.04, CADD 12.10
- H55Y (p.His55Tyr), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99786, Variant assessed as somatic; moderate impact.
- G56E (p.Gly56Glu), gnomAD rs1461624485, REVEL 0.05, CADD 7.88
- G56R (p.Gly56Arg), rs767419937, NCI-TCGA Cosmic COSV9978, cosmic curated COSV99786, REVEL 0.14, CADD 16.20, Variant assessed as somatic; moderate impact.
- G56W (p.Gly56Trp), cosmic curated COSV99784, REVEL 0.10, CADD 22.10
- G57D (p.Gly57Asp), gnomAD rs1760892116, REVEL 0.09, CADD 14.50
- G57S (p.Gly57Ser), gnomAD rs1167109152, CADD 0.59
- G58E (p.Gly58Glu), cosmic curated COSV55231
- G58R (p.Gly58Arg), cosmic curated COSV55228, TOPMed rs1206946298, gnomAD rs1206946298, REVEL 0.15, CADD 11.60
- G58V (p.Gly58Val), gnomAD rs1417757332, REVEL 0.20, CADD 15.10
- R59K (p.Arg59Lys), rs1257578125, NCI-TCGA Cosmic COSV5521, cosmic curated COSV55217, TOPMed rs1257578125, REVEL 0.10, AlphaMissense 0.13, Variant assessed as somatic; moderate impact.
- G61R (p.Gly61Arg), TOPMed rs1760891369, gnomAD rs1760891369, REVEL 0.02, CADD 17.80
- P62L (p.Pro62Leu), ESP rs377095820, ExAC rs377095820, TOPMed rs377095820, gnomAD rs377095820, REVEL 0.21, CADD 24.00, Uncertain significance, Inborn genetic diseases
- A63S (p.Ala63Ser), gnomAD rs1195602589, REVEL 0.03, AlphaMissense 0.08
- A63T (p.Ala63Thr), cosmic curated COSV55231, gnomAD rs1195602589, REVEL 0.04, AlphaMissense 0.07, Uncertain significance, Inborn genetic diseases
- A63V (p.Ala63Val), cosmic curated COSV55218, ExAC rs775327970, TOPMed rs775327970, gnomAD rs775327970, REVEL 0.04, AlphaMissense 0.17
- G64E (p.Gly64Glu), NCI-TCGA Cosmic COSV5521, cosmic curated COSV55215, REVEL 0.17, AlphaMissense 0.13, Variant assessed as somatic; moderate impact.
- G64R (p.Gly64Arg), TOPMed rs1360402468, gnomAD rs1360402468, CADD 9.41, Uncertain significance, Inborn genetic diseases
- T65N (p.Thr65Asn), gnomAD rs1211266501, REVEL 0.11, CADD 19.30
- S66L (p.Ser66Leu), TOPMed rs879654700, gnomAD rs879654700, REVEL 0.04, CADD 18.70
- G70A (p.Gly70Ala), gnomAD rs1305953474
- G70D (p.Gly70Asp), gnomAD rs1305953474, Uncertain significance, Inborn genetic diseases
- G70S (p.Gly70Ser), ExAC rs748637172, TOPMed rs748637172, gnomAD rs748637172
- G74A (p.Gly74Ala), gnomAD rs1328240186, REVEL 0.18, CADD 19.30
- G74E (p.Gly74Glu), cosmic curated COSV99786
- G74R (p.Gly74Arg), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99785, Variant assessed as somatic; moderate impact.
- G74V (p.Gly74Val), gnomAD rs1328240186, REVEL 0.24, CADD 23.50
- I75M (p.Ile75Met), cosmic curated COSV10960
- I75T (p.Ile75Thr), ExAC rs749499641, gnomAD rs749499641, REVEL 0.16, CADD 22.30, Uncertain significance, Inborn genetic diseases
- G76D (p.Gly76Asp), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- H78Q (p.His78Gln), TOPMed rs1760889132
- H78R (p.His78Arg), cosmic curated COSV10605
- A80P (p.Ala80Pro), Ensembl rs1760889058, CADD 1.45
- T83I (p.Thr83Ile), cosmic curated COSV10807
- T83K (p.Thr83Lys), TOPMed rs1027738394, gnomAD rs1027738394, REVEL 0.07, AlphaMissense 0.35
- T83R (p.Thr83Arg), TOPMed rs1027738394, gnomAD rs1027738394, REVEL 0.10, AlphaMissense 0.11
- G84E (p.Gly84Glu), ExAC rs780323436, gnomAD rs780323436, REVEL 0.20, CADD 19.00
- G84W (p.Gly84Trp), gnomAD rs1181535350, REVEL 0.23, CADD 23.40
- S88C (p.Ser88Cys), TOPMed rs1760888355, gnomAD rs1760888355, REVEL 0.27, AlphaMissense 0.08
- S88F (p.Ser88Phe), cosmic curated COSV10454
- P89L (p.Pro89Leu), TOPMed rs1191399862, gnomAD rs1191399862, REVEL 0.18, AlphaMissense 0.16, Uncertain significance, Inborn genetic diseases
- P89S (p.Pro89Ser), cosmic curated COSV55216
- P89T (p.Pro89Thr), cosmic curated COSV55230, REVEL 0.13, CADD 19.30
- P90L (p.Pro90Leu), 1000Genomes rs540296376, ExAC rs540296376, gnomAD rs540296376, REVEL 0.17, AlphaMissense 0.14
- P90S (p.Pro90Ser), Ensembl rs2113414490, REVEL 0.11, CADD 18.40
- S91G (p.Ser91Gly), ExAC rs763922754, gnomAD rs763922754, REVEL 0.10, CADD 19.70
- A92G (p.Ala92Gly), gnomAD rs1332659864, REVEL 0.12, AlphaMissense 0.61
- A92T (p.Ala92Thr), rs200659914, ClinGen CA3645673, cosmic curated COSV55211, ClinVar RCV002960643, CADD 9.83, Uncertain significance, Inborn genetic diseases
- P93S (p.Pro93Ser), cosmic curated COSV55228, gnomAD rs1301020086, REVEL 0.09, AlphaMissense 0.47
- P93T (p.Pro93Thr), cosmic curated COSV55231
- R94G (p.Arg94Gly), ESP rs142423255, ExAC rs142423255, TOPMed rs142423255, gnomAD rs142423255, REVEL 0.28, CADD 24.00
- R94M (p.Arg94Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- R94W (p.Arg94Trp), ESP rs142423255, ExAC rs142423255, TOPMed rs142423255, gnomAD rs142423255, REVEL 0.31, CADD 25.00
- S95F (p.Ser95Phe), cosmic curated COSV55223, TOPMed rs139030983, gnomAD rs139030983, REVEL 0.25, AlphaMissense 0.36
- V96I (p.Val96Ile), TOPMed rs1760886290, CADD 4.96
- P97H (p.Pro97His), gnomAD rs867470111, REVEL 0.35, AlphaMissense 0.18
- P97L (p.Pro97Leu), rs867470111, NCI-TCGA Cosmic COSV5522, cosmic curated COSV55222, gnomAD rs867470111, AlphaMissense 0.18, MetaLR 0.55, Variant assessed as somatic; moderate impact.
- P97S (p.Pro97Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V98M (p.Val98Met), cosmic curated COSV10807, ExAC rs765851071, gnomAD rs765851071, REVEL 0.05, AlphaMissense 0.73
- A99G (p.Ala99Gly), cosmic curated COSV10584, TOPMed rs1052847025, gnomAD rs1052847025, REVEL 0.10, AlphaMissense 0.16, Uncertain significance, Inborn genetic diseases
- A99V (p.Ala99Val), TOPMed rs1052847025, gnomAD rs1052847025, REVEL 0.09, AlphaMissense 0.26, Uncertain significance
- T100A (p.Thr100Ala), Ensembl rs904315425
- T101M (p.Thr101Met), 1000Genomes rs144411643, ESP rs144411643, ExAC rs144411643, TOPMed rs144411643, REVEL 0.21, AlphaMissense 0.69, Likely benign, ATXN1-related disorder
- P103S (p.Pro103Ser), TOPMed rs1237734956, gnomAD rs1237734956, REVEL 0.53, AlphaMissense 0.83
- A104V (p.Ala104Val), NCI-TCGA Cosmic COSV5520, cosmic curated COSV55207, REVEL 0.14, CADD 22.90, Variant assessed as somatic; moderate impact.
- A105P (p.Ala105Pro), cosmic curated COSV55212, 1000Genomes rs150050637, ESP rs150050637, ExAC rs150050637, REVEL 0.08, AlphaMissense 0.31
- A105T (p.Ala105Thr), cosmic curated COSV55212, 1000Genomes rs150050637, ESP rs150050637, ExAC rs150050637, REVEL 0.03, AlphaMissense 0.10
- A105V (p.Ala105Val), cosmic curated COSV55229, ExAC rs781297445, TOPMed rs781297445, gnomAD rs781297445, REVEL 0.12, AlphaMissense 0.19, Likely benign, Inborn genetic diseases
- Y106C (p.Tyr106Cys), ExAC rs746951702, gnomAD rs746951702, REVEL 0.26, AlphaMissense 0.06
- A107T (p.Ala107Thr), ExAC rs758412921, TOPMed rs758412921, gnomAD rs758412921, REVEL 0.18, CADD 13.30, Uncertain significance, Inborn genetic diseases
- A107V (p.Ala107Val), rs1333234060, NCI-TCGA Cosmic COSV5520, cosmic curated COSV55208, Ensembl rs1333234060, AlphaMissense 0.09, MetaLR 0.16, Variant assessed as somatic; moderate impact.
- T108I (p.Thr108Ile), Ensembl rs1760883557, REVEL 0.24, CADD 19.30
- P109A (p.Pro109Ala), TOPMed rs1035345633, gnomAD rs1035345633, REVEL 0.18, CADD 12.40
- P109L (p.Pro109Leu), rs752493191, NCI-TCGA Cosmic COSV5522, cosmic curated COSV55228, ExAC rs752493191, REVEL 0.40, CADD 23.10, Variant assessed as somatic; moderate impact.
- G112V (p.Gly112Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- T113I (p.Thr113Ile), ESP rs367700814, TOPMed rs367700814, gnomAD rs367700814, REVEL 0.18, AlphaMissense 0.09
- T113N (p.Thr113Asn), ESP rs367700814, TOPMed rs367700814, gnomAD rs367700814
- P114L (p.Pro114Leu), TOPMed rs1397068418, gnomAD rs1397068418, REVEL 0.21, AlphaMissense 0.10
- P114S (p.Pro114Ser), TOPMed rs866720611
- V115G (p.Val115Gly), gnomAD rs1318043784
- V115L (p.Val115Leu), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99787, Variant assessed as somatic; moderate impact.
- S116Y (p.Ser116Tyr), TOPMed rs1166684970, REVEL 0.52, CADD 25.60
- V118L (p.Val118Leu), cosmic curated COSV55222
- V118M (p.Val118Met), rs1390386736, NCI-TCGA Cosmic COSV5522, NCI-TCGA Cosmic COSV9978, cosmic curated COSV99787, REVEL 0.30, AlphaMissense 0.07, Variant assessed as somatic; moderate impact.
- Q119R (p.Gln119Arg), 1000Genomes rs567297318, ExAC rs567297318, TOPMed rs567297318, gnomAD rs567297318, REVEL 0.56, AlphaMissense 0.11, Uncertain significance, Inborn genetic diseases
- Y120C (p.Tyr120Cys), NCI-TCGA Cosmic COSV5522, cosmic curated COSV55228, Variant assessed as somatic; moderate impact.
- Y120H (p.Tyr120His), rs763470838, ExAC rs763470838, gnomAD rs763470838, REVEL 0.73, CADD 27.00, Variant assessed as somatic; moderate impact.
- A121S (p.Ala121Ser), ExAC rs770179993, gnomAD rs770179993, REVEL 0.20, CADD 18.90
- A121T (p.Ala121Thr), rs770179993, cosmic curated COSV10807, ExAC rs770179993, gnomAD rs770179993, REVEL 0.16, CADD 13.20, Variant assessed as somatic; moderate impact.
- A121V (p.Ala121Val), gnomAD rs1760880466, REVEL 0.38, CADD 24.10
- L123R (p.Leu123Arg), NCI-TCGA Cosmic COSV5521, cosmic curated COSV55213, Variant assessed as somatic; moderate impact.
- P124L (p.Pro124Leu), gnomAD rs1255400842, REVEL 0.25, CADD 23.30
- H125R (p.His125Arg), gnomAD rs1483290144
- T126P (p.Thr126Pro), Ensembl rs1581692663
- F127C (p.Phe127Cys), ExAC rs776775767, gnomAD rs776775767, REVEL 0.34, CADD 24.50
- I130L (p.Ile130Leu), ESP rs147449173, ExAC rs147449173, TOPMed rs147449173, gnomAD rs147449173, REVEL 0.13, CADD 23.40, Uncertain significance, Inborn genetic diseases
- I130S (p.Ile130Ser), ExAC rs746993452, TOPMed rs746993452, gnomAD rs746993452, REVEL 0.32, CADD 26.70
- I130T (p.Ile130Thr), ExAC rs746993452, TOPMed rs746993452, gnomAD rs746993452, REVEL 0.30, CADD 25.40
- G131E (p.Gly131Glu), ExAC rs772096581
- S132Y (p.Ser132Tyr), TOPMed rs1760878739
- S133F (p.Ser133Phe), NCI-TCGA TCGA novel, REVEL 0.26, CADD 26.60, Variant assessed as somatic; moderate impact.
- Q134* (p.Gln134Ter), Ensembl rs1760878327
- Q134L (p.Gln134Leu), NCI-TCGA Cosmic COSV9978, cosmic curated COSV99785, Variant assessed as somatic; moderate impact.
- Y135* (p.Tyr135Ter), NCI-TCGA Cosmic COSV5521, cosmic curated COSV55215, Variant assessed as somatic; high impact.
- Y135C (p.Tyr135Cys), TOPMed rs1760878079, REVEL 0.33, AlphaMissense 0.15
Public ATXN1 analysis runs
- ATXN1 analysis run — ATXN1 (1,547 variants) — completed 2026-08-22