ATP6V1B1 (P15313) variants and mutations
ATP6V1B1 (also known as P15313) is a human protein-coding gene encoding a v-type proton ATPase subunit B, kidney isoform protein. It supplies an essential catalytic subunit of the vacuolar proton pump in acid-secreting epithelia, including renal intercalated cells and the inner ear. Biallelic loss-of-function variants cause distal renal tubular acidosis, often accompanied by sensorineural hearing loss. This analysis covers 861 ATP6V1B1 variants and mutations. Of these, 78% have computational variant effect predictions. Disease context includes renal tubular acidosis, distal, 2, with progressive sensorineural hearing loss, distal renal tubular acidosis, and hereditary disease. Example ATP6V1B1 variants include M1L, M1T, and A2D.
Variant analysis overview
- Gene: ATP6V1B1
- Protein: P15313
- UniProt accession: P15313
- Organism: Homo sapiens
- Variants analyzed: 861
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 687 unspecified-consequence records; 67 synonymous variants; 21 frameshift variants; 76 missense variants; 3 stop-gained variants; 5 splice-region variants; 3 substitution
- Prediction scores: 668 variants have prediction scores (78% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: renal tubular acidosis, distal, 2, with progressive sensorineural hearing loss, distal renal tubular acidosis, hereditary disease, nephrocalcinosis, autosomal recessive distal renal tubular acidosis, polydactyly, postaxial, type A1, Rare genetic deafness, renal tubular acidosis, gout, renal tubular acidosis, distal, 3, with or without sensorineural hearing loss, disease of genitourinary system, urogenital tract malformation.
Protein structure and variant hotspots
- Protein features: 1 binding sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable ATP6V1B1 variants
Examples include M1L, M1T, A2D, A2S, A2T, A2V, A2A, M3T. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1L (p.Met1Leu), rs1553415231, ClinGen CA347176656, ClinVar RCV001230448, ClinVar RCV002491738, MetaLR 0.39, MetaSVM -0.49, Uncertain significance, not provided; Renal tubular acidosis with progressive nerve deafness
- M1T (p.Met1Thr), rs11681642, ClinGen CA133784, ClinVar RCV000037207, ClinVar RCV000345623, MetaLR 0.00, MetaSVM -1.08, Benign, not specified; not provided; Renal tubular acidosis with progressive nerve deafn
- A2D (p.Ala2Asp), rs876657744, ClinGen CA10577204, ClinVar RCV000219935, ClinVar RCV001833188, REVEL 0.36, CADD 24.10, Uncertain significance, not specified
- A2S (p.Ala2Ser), rs142881463, ClinGen CA1700808, ClinVar RCV001581479, ClinVar RCV001836456, REVEL 0.28, CADD 24.40, Uncertain significance, Inborn genetic diseases; not provided; Renal tubular acidosis with progressive n
- A2T (p.Ala2Thr), ESP rs142881463, ExAC rs142881463, TOPMed rs142881463, gnomAD rs142881463, Uncertain significance
- A2V (p.Ala2Val), NCI-TCGA Cosmic COSV5226, cosmic curated COSV52266, Variant assessed as somatic; moderate impact.
- A2A (p.Ala2Ala), rs1553415239, gnomAD 2-70935960-C-G, CADD 8.89
- M3T (p.Met3Thr), ExAC rs782330616, TOPMed rs782330616, gnomAD rs782330616, REVEL 0.23, CADD 1.88
- M3V (p.Met3Val), TOPMed rs1444142592, REVEL 0.24, CADD 5.69
- E4G (p.Glu4Gly), rs781974215, gnomAD 2-70935961-ATGGAG, CADD 26.70
- E4K (p.Glu4Lys), gnomAD 2-70935964-G-A, REVEL 0.19, CADD 5.07
- I5M (p.Ile5Met), NCI-TCGA Cosmic COSV9931, cosmic curated COSV99313, REVEL 0.20, CADD 20.10, Uncertain significance, Renal tubular acidosis with progressive nerve deafness
- I5T (p.Ile5Thr), TOPMed rs1679840359, REVEL 0.22, CADD 22.70
- D6E (p.Asp6Glu), rs2104795225, ClinGen CA347176697, ClinVar RCV002462724, REVEL 0.18, CADD 16.60, Uncertain significance, not provided
- D6A (p.Asp6Ala), gnomAD 2-70935968-TAGAC-, CADD 27.80
- D6D (p.Asp6Asp), rs2104795225, gnomAD 2-70935972-C-T, CADD 10.10
- S7S (p.Ser7Ser), gnomAD 2-70935975-C-T, CADD 7.72
- R8M (p.Arg8Met), TOPMed rs1553415242, gnomAD rs1553415242, REVEL 0.41, CADD 22.20
- R8R (p.Arg8Arg), gnomAD 2-70935976-A-C, CADD 9.39
- R8K (p.Arg8Lys), gnomAD 2-70935977-G-A, REVEL 0.31, CADD 20.70
- P9H (p.Pro9His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P9S (p.Pro9Ser), NCI-TCGA Cosmic COSV5226, cosmic curated COSV52265, REVEL 0.24, CADD 3.46, Variant assessed as somatic; moderate impact.
- P9T (p.Pro9Thr), Ensembl rs1679840462, REVEL 0.18, CADD 8.72
- P9P (p.Pro9Pro), rs17853498, gnomAD 2-70935981-T-C, CADD 3.90
- G10A (p.Gly10Ala), TOPMed rs879967148, gnomAD rs879967148, REVEL 0.23, CADD 11.20
- G10E (p.Gly10Glu), TOPMed rs879967148, gnomAD rs879967148, REVEL 0.25, CADD 12.80
- G10R (p.Gly10Arg), ExAC rs782237301, TOPMed rs782237301, gnomAD rs782237301, REVEL 0.17, CADD 11.40
- G10V (p.Gly10Val), TOPMed rs879967148, gnomAD rs879967148, REVEL 0.16, CADD 12.50, Uncertain significance, Inborn genetic diseases
- G10W (p.Gly10Trp), rs2104795239, gnomAD 2-70935978-G-GC, CADD 23.20
- G10G (p.Gly10Gly), rs782382032, gnomAD 2-70935984-G-C, CADD 4.55
- G11E (p.Gly11Glu), TOPMed rs1053770030, gnomAD rs1053770030, REVEL 0.14, CADD 15.00, Uncertain significance, Inborn genetic diseases
- G11R (p.Gly11Arg), ExAC rs781992150, TOPMed rs781992150, gnomAD rs781992150, REVEL 0.14, CADD 17.40, Uncertain significance, Renal tubular acidosis with progressive nerve deafness
- G11W (p.Gly11Trp), gnomAD 2-70935985-G-T, REVEL 0.35, CADD 22.60
- G11G (p.Gly11Gly), rs199559744, gnomAD 2-70935987-G-A, CADD 1.79
- L12F (p.Leu12Phe), NCI-TCGA Cosmic COSV5226, NCI-TCGA Cosmic COSV9931, cosmic curated COSV99313, Variant assessed as somatic; moderate impact.
- L12S (p.Leu12Ser), rs782052865, gnomAD 2-70935980-CT-C, CADD 13.40
- L12A (p.Leu12Ala), rs1679840748, gnomAD 2-70935981-T-TG, CADD 22.30
- L12L (p.Leu12Leu), rs781923112, gnomAD 2-70935990-C-A, CADD 5.25
- P13S (p.Pro13Ser), gnomAD rs1553415256
- P13P (p.Pro13Pro), rs782066627, gnomAD 2-70935993-C-T, CADD 0.62
- G14A (p.Gly14Ala), rs782513986, ClinGen CA49687422, ClinVar RCV003210084, ClinVar RCV005029939, REVEL 0.22, CADD 12.40, Uncertain significance, Inborn genetic diseases; Renal tubular acidosis with progressive nerve deafness
- G14R (p.Gly14Arg), rs111306070, ClinGen CA1700820, ClinVar RCV002855969, 1000Genomes rs111306070, REVEL 0.30, CADD 0.01, Uncertain significance, Inborn genetic diseases
- G14S (p.Gly14Ser), rs111306070, ClinGen CA1700819, ClinVar RCV000939451, ClinVar RCV001137237, REVEL 0.28, CADD 0.00, Benign/Likely benign, not specified; not provided; Renal tubular acidosis with progressive nerve deafn
- G14G (p.Gly14Gly), gnomAD 2-70935996-C-T, CADD 7.30
- S15N (p.Ser15Asn), gnomAD 2-70935998-G-A, REVEL 0.10, CADD 2.78
- S15S (p.Ser15Ser), rs1045132687, gnomAD 2-70935999-T-C, CADD 3.28
- S16G (p.Ser16Gly), Ensembl rs2104795299
- S16R (p.Ser16Arg), gnomAD rs1553415265, REVEL 0.13, CADD 5.95
- S16T (p.Ser16Thr), 1000Genomes rs552163310, ExAC rs552163310, gnomAD rs552163310, REVEL 0.12, CADD 0.20
- C17Y (p.Cys17Tyr), rs782793493, ExAC rs782793493, TOPMed rs782793493, gnomAD rs782793493, REVEL 0.16, CADD 8.73, Variant assessed as somatic; moderate impact.
- N18S (p.Asn18Ser), Ensembl rs1679841572, REVEL 0.10, CADD 4.69, Uncertain significance, Inborn genetic diseases
- N18H (p.Asn18His), gnomAD 2-70936006-A-C, REVEL 0.12, CADD 7.34
- L19* (p.Leu19Ter), gnomAD 2-70936007-AC-A, CADD 14.90
- G20A (p.Gly20Ala), cosmic curated COSV99313, TOPMed rs1418218970, gnomAD rs1418218970, REVEL 0.21, AlphaMissense 0.06
- G20R (p.Gly20Arg), Ensembl rs1558666367
- G20V (p.Gly20Val), rs1418218970, NCI-TCGA Cosmic COSV9931, cosmic curated COSV99313, AlphaMissense 0.06, MetaLR 0.19, Variant assessed as somatic; moderate impact.
- G20D (p.Gly20Asp), gnomAD 2-70936013-G-A, REVEL 0.44, CADD 11.20
- G20G (p.Gly20Gly), rs1679841739, gnomAD 2-70936014-T-G, CADD 2.98
- A21T (p.Ala21Thr), gnomAD 2-70936015-G-A, REVEL 0.14, CADD 5.77
- A21S (p.Ala21Ser), gnomAD 2-70936015-G-T, REVEL 0.12, CADD 0.37
- A22P (p.Ala22Pro), Ensembl rs1679841825
- A22V (p.Ala22Val), 1000Genomes rs570549292, ExAC rs570549292, gnomAD rs570549292, REVEL 0.26, CADD 15.50
- R23* (p.Arg23Ter), rs1553415274, ClinGen CA347176795, NCI-TCGA Cosmic COSV5226, cosmic curated COSV52266, Pathogenic
- R23P (p.Arg23Pro), ExAC rs782447716, TOPMed rs782447716, gnomAD rs782447716, REVEL 0.58, CADD 14.60, Uncertain significance
- R23Q (p.Arg23Gln), rs782447716, ClinGen CA347176796, ClinVar RCV002793557, ClinVar RCV005028364, REVEL 0.16, CADD 7.59, Uncertain significance, Renal tubular acidosis with progressive nerve deafness; Inborn genetic diseases
- R23G (p.Arg23Gly), gnomAD 2-70936021-C-G, REVEL 0.43, CADD 14.90
- R23R (p.Arg23Arg), rs1473102623, gnomAD 2-70936023-A-G, CADD 2.40
- E24* (p.Glu24Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- E24R (p.Glu24Arg), rs1405534436, gnomAD 2-70936021-C-CG, CADD 18.40
- E24E (p.Glu24Glu), rs782572595, gnomAD 2-70936026-A-G, CADD 4.31
- H25H (p.His25His), rs782596977, gnomAD 2-70936029-C-T, CADD 3.92
- M26I (p.Met26Ile), ExAC rs782635244, gnomAD rs782635244, REVEL 0.15, CADD 15.70
- M26T (p.Met26Thr), rs527738649, ClinGen CA1700827, ClinVar RCV000222331, ClinVar RCV000766323, REVEL 0.14, CADD 14.60, Conflicting interpretations, not provided; not specified
- M26V (p.Met26Val), rs781815747, ClinGen CA1700826, ClinVar RCV002976301, ClinVar RCV003367929, REVEL 0.13, CADD 0.00, Conflicting interpretations, Inborn genetic diseases; not provided
- M26R (p.Met26Arg), gnomAD 2-70936031-T-G, REVEL 0.21, CADD 16.40
- Q27* (p.Gln27Ter), rs1288346981, ClinGen CA347176822, ClinVar RCV001328240, ClinVar RCV003558784, CADD 41.00, Pathogenic
- Q27E (p.Gln27Glu), gnomAD 2-70936033-C-G, REVEL 0.20, CADD 15.50
- Q27Q (p.Gln27Gln), rs782255641, gnomAD 2-70936035-G-A, CADD 8.97
- A28E (p.Ala28Glu), 1000Genomes rs200569195, ExAC rs200569195, gnomAD rs200569195, REVEL 0.64, CADD 23.80, Uncertain significance, Renal tubular acidosis with progressive nerve deafness
- A28V (p.Ala28Val), rs200569195, ClinGen CA1700830, cosmic curated COSV52267, ClinVar RCV004418756, REVEL 0.47, CADD 24.30, Uncertain significance, not provided; Inborn genetic diseases
- A28P (p.Ala28Pro), gnomAD 2-70936036-G-C, REVEL 0.71, CADD 26.40
- A28G (p.Ala28Gly), gnomAD 2-70936037-C-G, REVEL 0.54, CADD 24.30
- A28A (p.Ala28Ala), rs374746874, gnomAD 2-70936038-G-A, CADD 8.22
- V29F (p.Val29Phe), gnomAD rs1553415284, REVEL 0.69, CADD 23.10
- V29I (p.Val29Ile), gnomAD rs1553415284
- T30I (p.Thr30Ile), rs17720303, ClinGen CA133790, cosmic curated COSV52265, ClinVar RCV000037210, REVEL 0.20, CADD 19.80, Benign/Likely benign, not specified; not provided; Renal tubular acidosis with progressive nerve deafn
- R31Q (p.Arg31Gln), rs143516810, cosmic curated COSV52265, ESP rs143516810, ExAC rs143516810, REVEL 0.41, CADD 23.50, Uncertain significance, Renal tubular acidosis with progressive nerve deafness
- R31R (p.Arg31Arg), rs121964879, gnomAD 2-70936045-C-A, CADD 10.10
- R31* (p.Arg31Ter), rs121964879, gnomAD 2-70936045-C-T, CADD 38.00
- N32K (p.Asn32Lys), NCI-TCGA Cosmic COSV5226, Variant assessed as somatic; moderate impact.
- N32S (p.Asn32Ser), gnomAD rs1553415290, REVEL 0.20, CADD 22.00
- N32T (p.Asn32Thr), gnomAD 2-70936046-GA-G, CADD 21.80
- N32N (p.Asn32Asn), rs2104795415, gnomAD 2-70936050-C-T, CADD 11.30
- Y33* (p.Tyr33Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- Y33N (p.Tyr33Asn), gnomAD 2-70936051-T-A, REVEL 0.79, CADD 26.20
- Y33Y (p.Tyr33Tyr), rs2104795418, gnomAD 2-70936053-C-T, CADD 9.34
- I34T (p.Ile34Thr), ExAC rs782229065, REVEL 0.44, CADD 22.00
- I34V (p.Ile34Val), gnomAD rs1553415291, REVEL 0.18, CADD 18.80
- I34N (p.Ile34Asn), gnomAD 2-70936055-T-A, REVEL 0.40, CADD 22.50
- T35N (p.Thr35Asn), cosmic curated COSV99029, TOPMed rs1015896794, gnomAD rs1015896794, REVEL 0.32, CADD 22.90, Uncertain significance, Inborn genetic diseases; Renal tubular acidosis with progressive nerve deafness
- T35P (p.Thr35Pro), Ensembl rs1572903344
- T35I (p.Thr35Ile), gnomAD 2-70936058-C-T, REVEL 0.42, CADD 20.60
- T35T (p.Thr35Thr), gnomAD 2-70936059-C-A, CADD 9.69
- H36P (p.His36Pro), Ensembl rs1572903350, REVEL 0.46, CADD 22.30
- H36Q (p.His36Gln), TOPMed rs1356717545, REVEL 0.12, CADD 13.10
- H36Y (p.His36Tyr), gnomAD 2-70936060-C-T, REVEL 0.43, CADD 22.90
- H36R (p.His36Arg), gnomAD 2-70936061-A-G, REVEL 0.15, CADD 20.40
- P37A (p.Pro37Ala), ExAC rs782369259, TOPMed rs782369259, gnomAD rs782369259, REVEL 0.50, CADD 22.80, Uncertain significance, Renal tubular acidosis with progressive nerve deafness
- P37S (p.Pro37Ser), gnomAD 2-70936063-C-T, REVEL 0.61, CADD 24.90
- P37L (p.Pro37Leu), gnomAD 2-70936064-C-T, REVEL 0.74, CADD 25.60
- P37H (p.Pro37His), gnomAD 2-70936064-C-A, REVEL 0.63, CADD 25.30
- P37R (p.Pro37Arg), gnomAD 2-70936064-C-G, REVEL 0.63, CADD 25.30
- P37P (p.Pro37Pro), gnomAD 2-70936065-C-G, CADD 9.91
- R38C (p.Arg38Cys), rs145773738, ClinGen CA1700836, cosmic curated COSV52265, ClinVar RCV001137239, REVEL 0.74, CADD 27.00, Uncertain significance, not provided; Renal tubular acidosis with progressive nerve deafness; ATP6V1B1-r
- R38H (p.Arg38His), rs782166295, ClinGen CA1700837, NCI-TCGA Cosmic COSV5226, cosmic curated COSV52267, REVEL 0.60, CADD 29.30, Uncertain significance, Inborn genetic diseases; not provided; Renal tubular acidosis with progressive n
- R38S (p.Arg38Ser), ESP rs145773738, ExAC rs145773738, TOPMed rs145773738, gnomAD rs145773738, REVEL 0.64, CADD 23.40, Uncertain significance
- R38P (p.Arg38Pro), rs1679843325, gnomAD 2-70936061-A-AC, CADD 27.80
- R38G (p.Arg38Gly), gnomAD 2-70936066-C-G, REVEL 0.65, CADD 23.50
- R38L (p.Arg38Leu), gnomAD 2-70936067-G-T, REVEL 0.67, CADD 23.40
- R38R (p.Arg38Arg), gnomAD 2-70936068-T-C, CADD 3.40
- T40S (p.Thr40Ser), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- T40T (p.Thr40Thr), gnomAD 2-70943659-C-T, CADD 13.60
- Y41* (p.Tyr41Ter), rs782151715, ClinGen CA347178458, ClinVar RCV002007589, ClinVar RCV005025515, CADD 39.00, Pathogenic
- Y41C (p.Tyr41Cys), NCI-TCGA Cosmic COSV5226, cosmic curated COSV52268, Variant assessed as somatic; moderate impact.
- Y41D (p.Tyr41Asp), ExAC rs782003525, gnomAD rs782003525
- Y41H (p.Tyr41His), ExAC rs782003525, gnomAD rs782003525, REVEL 0.82, CADD 26.50
- Y41Y (p.Tyr41Tyr), rs782151715, gnomAD 2-70943662-C-T, CADD 12.20
- R42G (p.Arg42Gly), Ensembl rs1680068412
- R42M (p.Arg42Met), gnomAD 2-70943664-G-T, REVEL 0.56, CADD 23.40
- R42K (p.Arg42Lys), gnomAD 2-70943664-G-A, REVEL 0.25, CADD 17.30
- R42S (p.Arg42Ser), gnomAD 2-70943665-G-T, REVEL 0.33, CADD 22.90
- R42R (p.Arg42Arg), rs782309945, gnomAD 2-70943665-G-A, CADD 10.90
- T43A (p.Thr43Ala), gnomAD rs1553416782, REVEL 0.61, CADD 23.80
- T43I (p.Thr43Ile), gnomAD rs1553416784, REVEL 0.60, CADD 22.60
- T43P (p.Thr43Pro), gnomAD 2-70943666-A-C, REVEL 0.80, CADD 25.00
- V44L (p.Val44Leu), rs781931952, ClinGen CA1700910, ClinVar RCV001864197, ExAC rs781931952, REVEL 0.63, CADD 22.10, Uncertain significance, not provided
- V44M (p.Val44Met), gnomAD 2-70943669-G-A, REVEL 0.72, CADD 25.70
- C45Y (p.Cys45Tyr), gnomAD rs1553416788, REVEL 0.59, CADD 22.50
- C45C (p.Cys45Cys), rs782078912, gnomAD 2-70943674-C-T, CADD 13.70
- S46G (p.Ser46Gly), ExAC rs782733702
- S46W (p.Ser46Trp), rs1553416787, gnomAD 2-70943670-TGTGCA, CADD 32.00
- S46S (p.Ser46Ser), rs2266918, gnomAD 2-70943677-C-T, CADD 4.04
- V47M (p.Val47Met), ExAC rs782128390, TOPMed rs782128390, gnomAD rs782128390, REVEL 0.81, CADD 24.90
- N48K (p.Asn48Lys), 1000Genomes rs144845223, ESP rs144845223, ExAC rs144845223, TOPMed rs144845223, REVEL 0.36, CADD 7.28, Benign
- N48N (p.Asn48Asn), rs144845223, gnomAD 2-70943683-C-T, CADD 1.86
- G49E (p.Gly49Glu), gnomAD rs1553416796, REVEL 0.97, CADD 25.60
- G49R (p.Gly49Arg), rs369442690, ClinGen CA1700915, ClinVar RCV003002156, ClinVar RCV004753605, REVEL 0.97, CADD 26.20, Uncertain significance, not provided
- G49W (p.Gly49Trp), ESP rs369442690, ExAC rs369442690, TOPMed rs369442690, gnomAD rs369442690, REVEL 0.97, CADD 27.20, Uncertain significance
- G49A (p.Gly49Ala), gnomAD 2-70943685-G-C, REVEL 0.97, CADD 24.90
- G49G (p.Gly49Gly), gnomAD 2-70943686-G-C, CADD 8.12
- P50S (p.Pro50Ser), Ensembl rs746617256, REVEL 0.73, CADD 24.50
- P50P (p.Pro50Pro), gnomAD 2-70943689-C-G, CADD 6.50
- L51M (p.Leu51Met), Ensembl rs1553416799
- L51G (p.Leu51Gly), gnomAD 2-70943686-GCC-G, CADD 26.40
- L51W (p.Leu51Trp), rs2104804994, gnomAD 2-70943686-GC-G, CADD 26.30
- L51L (p.Leu51Leu), gnomAD 2-70943692-G-A, CADD 10.60
- V52A (p.Val52Ala), NCI-TCGA Cosmic COSV5227, cosmic curated COSV52272, Variant assessed as somatic; moderate impact.
- V52L (p.Val52Leu), TOPMed rs1553416800, gnomAD rs1553416800, REVEL 0.71, CADD 22.00, Uncertain significance
- V52M (p.Val52Met), rs1553416800, TOPMed rs1553416800, gnomAD rs1553416800, REVEL 0.72, CADD 23.40, Uncertain significance, Inborn genetic diseases; Renal tubular acidosis with progressive nerve deafness
- V52V (p.Val52Val), gnomAD 2-70943695-G-A, CADD 9.82
- V53M (p.Val53Met), rs782734529, ClinGen CA1700916, ClinVar RCV002630086, ExAC rs782734529, REVEL 0.53, CADD 22.90, Uncertain significance, not provided
- V53A (p.Val53Ala), gnomAD 2-70943697-T-C, REVEL 0.59, CADD 22.90
- V53V (p.Val53Val), rs1361849084, gnomAD 2-70943698-G-T, CADD 8.34
- L54M (p.Leu54Met), TOPMed rs1267945831, gnomAD rs1267945831, REVEL 0.69, CADD 24.00
- L54P (p.Leu54Pro), TOPMed rs1680069838
- L54L (p.Leu54Leu), gnomAD 2-70943699-C-T, CADD 10.40
- L54R (p.Leu54Arg), gnomAD 2-70943700-T-G, REVEL 0.93, CADD 31.00
- D55Y (p.Asp55Tyr), gnomAD rs1553416804, REVEL 0.85, CADD 27.50
- D55N (p.Asp55Asn), gnomAD 2-70943702-G-A, REVEL 0.45, CADD 23.10
- D55G (p.Asp55Gly), gnomAD 2-70943703-A-G, REVEL 0.60, CADD 25.70
- D55A (p.Asp55Ala), gnomAD 2-70943703-A-C, REVEL 0.66, CADD 24.60
- R56G (p.Arg56Gly), rs781824659, ClinGen CA1700917, ClinVar RCV003070792, ExAC rs781824659, REVEL 0.33, CADD 20.60, Uncertain significance, not provided
- R56Q (p.Arg56Gln), rs782628302, ClinGen CA1700919, cosmic curated COSV10608, ClinVar RCV002011230, REVEL 0.25, CADD 18.60, Uncertain significance, not provided
- R56W (p.Arg56Trp), cosmic curated COSV52268, ExAC rs781824659, TOPMed rs781824659, gnomAD rs781824659, REVEL 0.43, CADD 26.80, Uncertain significance, not provided
- R56* (p.Arg56Ter), gnomAD 2-70943678-G-GTGA, CADD 25.70
- R56P (p.Arg56Pro), gnomAD 2-70943706-G-C, REVEL 0.48, CADD 22.70
- R56L (p.Arg56Leu), gnomAD 2-70943706-G-T, REVEL 0.33, CADD 20.20
- R56R (p.Arg56Arg), rs1438456940, gnomAD 2-70943707-G-C, CADD 7.64
- V57A (p.Val57Ala), gnomAD rs1553416809, REVEL 0.76, CADD 23.70
- V57I (p.Val57Ile), TOPMed rs1355993805, gnomAD rs1355993805, REVEL 0.47, CADD 21.90
Public ATP6V1B1 analysis runs
- ATP6V1B1 analysis run — ATP6V1B1 (861 variants) — completed 2026-08-21