ATP1A2 (P50993) variants and mutations
ATP1A2 (also known as P50993) is a human protein-coding gene encoding a sodium/potassium-transporting ATPase subunit alpha-2 protein. It restores sodium and potassium gradients after activity in astrocytes and other excitable tissues and thereby supports neuronal ion homeostasis. Pathogenic variants are a major cause of familial hemiplegic migraine type 2 and can produce severe episodic neurologic disease. This analysis covers 1,218 ATP1A2 variants and mutations. Of these, 69% have computational variant effect predictions. Disease context includes migraine, familial hemiplegic, 2, alternating hemiplegia of childhood 1, and developmental and epileptic encephalopathy 98. Example ATP1A2 variants include M1?, M1T, and G2C.
Variant analysis overview
- Gene: ATP1A2
- Protein: P50993
- UniProt accession: P50993
- Organism: Homo sapiens
- Variants analyzed: 1218
- Variant scope: all variants
- Completed: 2026-08-18
Variant and mutation evidence
- Variant composition: 1,054 unspecified-consequence records; 70 missense variants; 73 synonymous variants; 4 splice-region variants; 5 stop-gained variants; 8 frameshift variants; 1 in-frame insertions; 1 in-frame deletions; 2 substitution
- Prediction scores: 838 variants have prediction scores (69% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: migraine, familial hemiplegic, 2, alternating hemiplegia of childhood 1, developmental and epileptic encephalopathy 98, fetal akinesia, respiratory insufficiency, microcephaly, polymicrogyria, and dys, alternating hemiplegia of childhood, familial or sporadic hemiplegic migraine, familial hemiplegic migraine, congestive heart failure, atrial fibrillation, heart failure, cardiovascular disorder, hereditary disease.
Protein structure and variant hotspots
- Protein features: 10 transmembrane segments; 4 binding sites; 10 post-translational modification sites.
- Structural context: 193 variants have structural context.
- PTM context: 16 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable ATP1A2 variants
Examples include M1?, M1T, G2C, G2V, G2G, R3C, R3H, R3S. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1?, NCI-TCGA Cosmic COSV1007, cosmic curated COSV10076, Variant assessed as somatic; high impact.
- M1T (p.Met1Thr), rs1651158379, ClinGen CA343224879, ClinVar RCV001323788, MetaLR 0.58, MetaSVM 0.19, Uncertain significance, Familial hemiplegic migraine
- G2C (p.Gly2Cys), gnomAD 1-160115865-G-T, REVEL 0.53, CADD 27.80
- G2V (p.Gly2Val), gnomAD 1-160115866-G-T, REVEL 0.55, CADD 24.20
- G2G (p.Gly2Gly), gnomAD 1-160115867-C-A, CADD 11.90
- R3C (p.Arg3Cys), rs755450946, ClinGen CA343224913, ClinVar RCV002016314, ClinVar RCV005250231, REVEL 0.44, CADD 23.70, Uncertain significance, not provided; Familial hemiplegic migraine
- R3H (p.Arg3His), rs781687346, ClinGen CA313325, cosmic curated COSV63404, ClinVar RCV000186804, REVEL 0.43, CADD 22.70, Conflicting interpretations, Familial hemiplegic migraine; not specified; not provided
- R3S (p.Arg3Ser), ExAC rs755450946, gnomAD rs755450946, REVEL 0.48, CADD 22.50, Uncertain significance
- R3P (p.Arg3Pro), gnomAD 1-160115869-G-C, REVEL 0.51, CADD 23.30
- R3L (p.Arg3Leu), gnomAD 1-160115869-G-T, REVEL 0.48, CADD 22.60
- G4R (p.Gly4Arg), rs2524837514, ClinGen CA343224936, ClinVar RCV002622652, Uncertain significance, Familial hemiplegic migraine
- G4W (p.Gly4Trp), gnomAD 1-160115871-G-T, REVEL 0.56, CADD 33.00
- G4V (p.Gly4Val), gnomAD 1-160115872-G-T, REVEL 0.43, CADD 23.80
- G4E (p.Gly4Glu), gnomAD 1-160115872-G-A, REVEL 0.43, CADD 23.30
- G4G (p.Gly4Gly), gnomAD 1-160115873-G-A, CADD 23.40
- A5D (p.Ala5Asp), Ensembl rs1651373455, REVEL 0.30, CADD 0.77
- A5S (p.Ala5Ser), rs776180843, ClinGen CA1194072, ClinVar RCV003030380, ExAC rs776180843, REVEL 0.24, CADD 18.50, Uncertain significance, Familial hemiplegic migraine
- A5T (p.Ala5Thr), gnomAD 1-160120906-G-A, REVEL 0.24, CADD 16.60
- G6C (p.Gly6Cys), gnomAD 1-160120909-G-T, REVEL 0.55, CADD 25.20
- G6S (p.Gly6Ser), gnomAD 1-160120909-G-A, REVEL 0.39, CADD 21.70
- G6V (p.Gly6Val), gnomAD 1-160120910-G-T, REVEL 0.47, CADD 24.00
- G6G (p.Gly6Gly), gnomAD 1-160120911-C-G, CADD 4.19
- R7C (p.Arg7Cys), rs761260548, ClinGen CA1194073, ClinVar RCV000716397, ClinVar RCV002312780, REVEL 0.49, AlphaMissense 0.15, Uncertain significance, Inborn genetic diseases; Familial hemiplegic migraine
- R7G (p.Arg7Gly), rs761260548, ClinGen CA343226909, ClinVar RCV001058781, ExAC rs761260548, AlphaMissense 0.15, MetaLR 0.54, Uncertain significance, Familial hemiplegic migraine
- R7H (p.Arg7His), rs764755889, ClinGen CA1194074, ClinVar RCV001968452, ClinVar RCV003238886, REVEL 0.33, AlphaMissense 0.28, Uncertain significance, Familial hemiplegic migraine; not provided
- R7P (p.Arg7Pro), rs764755889, ClinGen CA343226917, ClinVar RCV002045520, ExAC rs764755889, AlphaMissense 0.28, MetaLR 0.60, Uncertain significance, Familial hemiplegic migraine
- R7S (p.Arg7Ser), gnomAD 1-160120912-C-A, REVEL 0.49, CADD 18.70
- R7L (p.Arg7Leu), gnomAD 1-160120913-G-T, REVEL 0.54, CADD 23.30
- R7R (p.Arg7Arg), gnomAD 1-160120914-T-C, CADD 0.32
- E8K (p.Glu8Lys), gnomAD rs1469623974, REVEL 0.30, CADD 22.10
- E8* (p.Glu8Ter), gnomAD 1-160120915-G-T, CADD 37.00
- E8Q (p.Glu8Gln), gnomAD 1-160120915-G-C, REVEL 0.21, CADD 20.00
- E8D (p.Glu8Asp), gnomAD 1-160120917-G-T, REVEL 0.29, CADD 14.50
- E8E (p.Glu8Glu), rs1651373826, gnomAD 1-160120917-G-A, CADD 7.55
- Y9N (p.Tyr9Asn), rs55858252, ClinGen CA313264, ClinVar RCV000186782, ClinVar RCV000229197, REVEL 0.28, CADD 21.30, Conflicting interpretations, Inborn genetic diseases; Fetal akinesia, respiratory insufficiency, microcephaly
- S10L (p.Ser10Leu), rs762611119, ClinGen CA1194075, ClinVar RCV000498736, ClinVar RCV006327103, REVEL 0.24, CADD 19.20, Uncertain significance, not provided; Inborn genetic diseases
- S10P (p.Ser10Pro), gnomAD 1-160120921-T-C, REVEL 0.33, CADD 20.30
- S10T (p.Ser10Thr), gnomAD 1-160120921-T-A, REVEL 0.19, CADD 15.80
- S10Y (p.Ser10Tyr), gnomAD 1-160120921-TC-T, CADD 24.40
- S10* (p.Ser10Ter), gnomAD 1-160120922-C-A, CADD 36.00
- P11S (p.Pro11Ser), TOPMed rs1432353546, gnomAD rs1432353546, REVEL 0.23, CADD 18.40, Uncertain significance, not provided
- P11T (p.Pro11Thr), gnomAD 1-160120924-C-A, REVEL 0.27, CADD 18.40
- P11H (p.Pro11His), gnomAD 1-160120925-C-A, REVEL 0.27, CADD 22.00
- P11P (p.Pro11Pro), gnomAD 1-160120926-T-A, CADD 7.61
- A12P (p.Ala12Pro), Ensembl rs2101983790
- A12V (p.Ala12Val), gnomAD 1-160120928-C-T, REVEL 0.31, CADD 20.20
- A12A (p.Ala12Ala), gnomAD 1-160120929-C-G, CADD 0.62
- A13S (p.Ala13Ser), ExAC rs753074130, TOPMed rs753074130, gnomAD rs753074130, REVEL 0.27, CADD 21.80, Uncertain significance
- A13T (p.Ala13Thr), rs753074130, ClinGen CA1194077, ClinVar RCV000517434, ClinVar RCV001364656, REVEL 0.23, CADD 22.50, Uncertain significance, Familial hemiplegic migraine; Inborn genetic diseases; not specified
- A13V (p.Ala13Val), rs1651374712, ClinGen CA343227100, ClinVar RCV003063936, ClinVar RCV005744591, REVEL 0.20, CADD 19.40, Uncertain significance, Inborn genetic diseases; Familial hemiplegic migraine
- p.Ala13dup, rs1172592755, gnomAD 1-160120926-T-TGC, CADD 17.40
- A13A (p.Ala13Ala), gnomAD 1-160120932-C-A, CADD 8.88
- T14I (p.Thr14Ile), gnomAD rs1327349113
- T14A (p.Thr14Ala), gnomAD 1-160120933-A-G, REVEL 0.19, CADD 16.10
- T14T (p.Thr14Thr), rs1335547839, gnomAD 1-160120935-C-T, CADD 8.61
- T15M (p.Thr15Met), rs371257019, ClinGen CA1194078, cosmic curated COSV10526, ClinVar RCV000430842, REVEL 0.21, CADD 20.30, Conflicting interpretations, Inborn genetic diseases; Familial hemiplegic migraine; not provided
- T15A (p.Thr15Ala), gnomAD 1-160120936-A-G, REVEL 0.24, CADD 18.80
- T15T (p.Thr15Thr), gnomAD 1-160120938-G-T, CADD 0.06
- A16T (p.Ala16Thr), rs754418656, ClinGen CA1194080, ClinVar RCV003118694, ExAC rs754418656, REVEL 0.17, CADD 10.30, Uncertain significance, Familial hemiplegic migraine
- A16S (p.Ala16Ser), gnomAD 1-160120939-G-T, REVEL 0.25, CADD 5.19
- A16E (p.Ala16Glu), gnomAD 1-160120940-C-A, REVEL 0.24, CADD 11.30
- A16V (p.Ala16Val), gnomAD 1-160120940-C-T, REVEL 0.24, CADD 17.40
- E17D (p.Glu17Asp), Ensembl rs1558002451, REVEL 0.27, CADD 14.40
- E17Q (p.Glu17Gln), gnomAD rs1233714976, REVEL 0.26, CADD 22.10
- E17* (p.Glu17Ter), gnomAD 1-160120942-G-T, CADD 38.00
- E17G (p.Glu17Gly), gnomAD 1-160120943-A-G, REVEL 0.23, CADD 23.30
- N18N (p.Asn18Asn), rs1281283645, gnomAD 1-160120947-T-C, CADD 11.80
- G19R (p.Gly19Arg), TOPMed rs1347478678, gnomAD rs1347478678, REVEL 0.33, CADD 22.70
- G19V (p.Gly19Val), rs757373744, ClinGen CA313319, ClinVar RCV000186802, ClinVar RCV005089934, REVEL 0.25, CADD 22.20, Uncertain significance, not provided; Familial hemiplegic migraine
- G19E (p.Gly19Glu), gnomAD 1-160120949-G-A, REVEL 0.25, CADD 21.00
- G19G (p.Gly19Gly), rs779140540, gnomAD 1-160120950-G-A, CADD 8.59
- G20D (p.Gly20Asp), rs1437032305, ClinGen CA343227273, ClinVar RCV001760933, gnomAD rs1437032305, REVEL 0.39, CADD 17.00, Uncertain significance, not provided
- G20S (p.Gly20Ser), rs1558002462, ClinGen CA343227251, ClinVar RCV000699400, Ensembl rs1558002462, AlphaMissense 0.08, MetaLR 0.47, Uncertain significance, Familial hemiplegic migraine
- G20A (p.Gly20Ala), gnomAD 1-160120947-TG-T, CADD 27.90
- G20G (p.Gly20Gly), rs746073352, gnomAD 1-160120953-C-T, CADD 6.24
- G21S (p.Gly21Ser), rs758613291, ClinGen CA1194083, ClinVar RCV001321305, ExAC rs758613291, REVEL 0.29, CADD 20.90, Likely benign, Familial hemiplegic migraine
- G21D (p.Gly21Asp), gnomAD 1-160120955-G-A, REVEL 0.33, CADD 21.60
- G21V (p.Gly21Val), gnomAD 1-160120955-G-T, REVEL 0.33, CADD 21.90
- K22N (p.Lys22Asn), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- K22K (p.Lys22Lys), gnomAD 1-160120959-G-A, CADD 11.80
- K23E (p.Lys23Glu), rs1651376133, ClinGen CA343227408, ClinVar RCV001070676, Ensembl rs1651376133, AlphaMissense 0.17, MetaLR 0.55, Uncertain significance, Familial hemiplegic migraine
- K23R (p.Lys23Arg), TOPMed rs1192524870, gnomAD rs1192524870, REVEL 0.16, CADD 22.60
- K23K (p.Lys23Lys), gnomAD 1-160120962-G-A, CADD 11.20
- Q25Q (p.Gln25Gln), rs2101983843, gnomAD 1-160120968-G-A, CADD 10.20
- Q25H (p.Gln25His), gnomAD 1-160120968-G-T, REVEL 0.32, CADD 22.70
- K26Q (p.Lys26Gln), Ensembl rs1651376405
- K26K (p.Lys26Lys), gnomAD 1-160120971-G-A, CADD 2.57
- E27D (p.Glu27Asp), NCI-TCGA Cosmic COSV6340, cosmic curated COSV63404, Variant assessed as somatic; moderate impact.
- E27K (p.Glu27Lys), gnomAD rs1443866755, REVEL 0.27, CADD 20.10, Uncertain significance, not provided
- E27V (p.Glu27Val), cosmic curated COSV10749, TOPMed rs1651376646, Uncertain significance, not provided
- E27del (p.Glu27del), gnomAD 1-160120969-AAGG-, CADD 19.50
- E27E (p.Glu27Glu), gnomAD 1-160120974-G-A, CADD 8.96
- K28M (p.Lys28Met), gnomAD rs1377838920, REVEL 0.45, CADD 23.40
- L30M (p.Leu30Met), gnomAD 1-160120981-C-A, REVEL 0.26, CADD 13.20
- D31N (p.Asp31Asn), rs779868172, ClinGen CA1194084, ClinVar RCV003747445, ExAC rs779868172, REVEL 0.35, CADD 23.80, Uncertain significance, Familial hemiplegic migraine
- D31E (p.Asp31Glu), gnomAD 1-160120986-T-A, REVEL 0.32, CADD 12.40
- D31D (p.Asp31Asp), rs1651376986, gnomAD 1-160120986-T-C, CADD 10.40
- E32E (p.Glu32Glu), rs746828144, gnomAD 1-160120989-G-A, CADD 10.40
- L33L (p.Leu33Leu), gnomAD 1-160120990-C-T, CADD 12.10
- K35K (p.Lys35Lys), gnomAD 1-160120998-G-A, CADD 12.50
- E36K (p.Glu36Lys), rs1651377160, ClinGen CA343228024, cosmic curated COSV63403, ClinVar RCV001222829, AlphaMissense 0.99, MetaLR 0.62, Uncertain significance, Familial hemiplegic migraine
- E36E (p.Glu36Glu), rs1553244021, gnomAD 1-160121001-G-A, CADD 8.15
- V37G (p.Val37Gly), gnomAD 1-160121002-GT-G, CADD 32.00
- V37V (p.Val37Val), gnomAD 1-160121004-G-T, CADD 8.88
- A38S (p.Ala38Ser), 1000Genomes rs201688946, ExAC rs201688946, TOPMed rs201688946, gnomAD rs201688946, REVEL 0.18, CADD 10.70, Uncertain significance, not provided
- A38T (p.Ala38Thr), rs201688946, ClinGen CA1194086, ClinVar RCV001226214, ClinVar RCV005909072, REVEL 0.15, CADD 16.30, Uncertain significance, Familial hemiplegic migraine
- M39I (p.Met39Ile), gnomAD rs1410907135
- M39T (p.Met39Thr), gnomAD 1-160121009-T-C, REVEL 0.37, CADD 20.80
- D40V (p.Asp40Val), gnomAD rs1327184824
- D41E (p.Asp41Glu), TOPMed rs1439633790, gnomAD rs1439633790, REVEL 0.28, CADD 17.30
- D41Y (p.Asp41Tyr), gnomAD 1-160121195-G-T, REVEL 0.75, CADD 26.40
- H42N (p.His42Asn), NCI-TCGA Cosmic COSV1007, cosmic curated COSV10076, Variant assessed as somatic; moderate impact.
- H42Y (p.His42Tyr), Ensembl rs1651384307
- H42H (p.His42His), rs750571104, gnomAD 1-160121200-C-T, CADD 11.20
- K43N (p.Lys43Asn), rs61734527, ClinGen CA343228460, ClinVar RCV002005663, 1000Genomes rs61734527, AlphaMissense 0.86, MetaLR 0.47, Uncertain significance, Familial hemiplegic migraine
- K43R (p.Lys43Arg), rs796052281, ClinGen CA313346, ClinVar RCV000186811, Ensembl rs796052281, REVEL 0.30, CADD 22.80, Uncertain significance, not provided
- K43K (p.Lys43Lys), rs61734527, gnomAD 1-160121203-G-A, AlphaMissense 0.86, MetaLR 0.47
- L44L (p.Leu44Leu), rs780086533, gnomAD 1-160121204-C-T, CADD 11.50
- S45P (p.Ser45Pro), Ensembl rs1651384906, Uncertain significance
- S45T (p.Ser45Thr), rs1651384906, ClinGen CA343228494, ClinVar RCV001351648, Ensembl rs1651384906, AlphaMissense 0.07, MetaLR 0.40, Uncertain significance, Familial hemiplegic migraine
- S45S (p.Ser45Ser), gnomAD 1-160121209-C-A, CADD 10.40
- L46L (p.Leu46Leu), gnomAD 1-160121210-T-C, CADD 9.95
- D47N (p.Asp47Asn), gnomAD 1-160121213-G-A, REVEL 0.46, CADD 25.10
- D47H (p.Asp47His), gnomAD 1-160121213-G-C, REVEL 0.60, CADD 29.70
- D47D (p.Asp47Asp), rs1327304211, gnomAD 1-160121215-T-C, CADD 10.30
- E48A (p.Glu48Ala), TOPMed rs1651385081
- E48D (p.Glu48Asp), NCI-TCGA Cosmic COSV1007, cosmic curated COSV10076, Variant assessed as somatic; moderate impact.
- E48Q (p.Glu48Gln), gnomAD 1-160121216-G-C, REVEL 0.57, CADD 23.80
- E48E (p.Glu48Glu), gnomAD 1-160121218-G-A, CADD 9.91
- L49V (p.Leu49Val), TOPMed rs1482264819
- G50D (p.Gly50Asp), NCI-TCGA TCGA novel, TOPMed rs1570983300, gnomAD rs1570983300, REVEL 0.31, CADD 18.80, Uncertain significance
- G50S (p.Gly50Ser), Ensembl rs1651385324
- G50V (p.Gly50Val), rs1570983300, ClinGen CA343228694, ClinVar RCV000818228, TOPMed rs1570983300, REVEL 0.31, CADD 17.00, Uncertain significance, Familial hemiplegic migraine
- G50A (p.Gly50Ala), rs1219005191, gnomAD 1-160121220-TG-T, CADD 23.90
- G50G (p.Gly50Gly), rs1294452603, gnomAD 1-160121224-C-A, CADD 8.43
- R51C (p.Arg51Cys), rs747283283, ClinGen CA1194101, NCI-TCGA Cosmic COSV6340, cosmic curated COSV63403, REVEL 0.53, CADD 23.10, Conflicting interpretations, Familial hemiplegic migraine; not provided; Migraine, familial hemiplegic, 2
- R51H (p.Arg51His), rs144106169, ClinGen CA1194102, ClinVar RCV000414480, ClinVar RCV000475103, REVEL 0.36, CADD 23.20, Conflicting interpretations, Familial hemiplegic migraine; not specified; Inborn genetic diseases
- R51L (p.Arg51Leu), rs144106169, ClinGen CA313322, ClinVar RCV000186803, ClinVar RCV001045545, REVEL 0.49, CADD 23.20, Uncertain significance, Familial hemiplegic migraine; not provided
- R51S (p.Arg51Ser), ExAC rs747283283, TOPMed rs747283283, gnomAD rs747283283, Benign
- R51G (p.Arg51Gly), gnomAD 1-160121225-C-G, REVEL 0.51, CADD 19.50
- K52I (p.Lys52Ile), NCI-TCGA Cosmic COSV6340, cosmic curated COSV63404, Variant assessed as somatic; moderate impact.
- Y53* (p.Tyr53Ter), ExAC rs748066442, TOPMed rs748066442, gnomAD rs748066442, CADD 36.00, Likely benign
- Y53C (p.Tyr53Cys), rs1651387702, ClinGen CA343228765, ClinVar RCV003061136, ClinVar RCV005233075, REVEL 0.85, CADD 28.40, Uncertain significance, Familial hemiplegic migraine; not provided
- Y53H (p.Tyr53His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- Y53W (p.Tyr53Trp), gnomAD 1-160121226-GCAAA, CADD 31.00
- Y53Y (p.Tyr53Tyr), rs748066442, gnomAD 1-160121233-C-T, CADD 7.14
- Q54* (p.Gln54Ter), NCI-TCGA Cosmic COSV6340, cosmic curated COSV63406, Variant assessed as somatic; high impact.
- Q54K (p.Gln54Lys), rs2524849489, ClinGen CA343228791, ClinVar RCV003746722, ClinVar RCV004723395, Uncertain significance, Familial hemiplegic migraine; Developmental and epileptic encephalopathy 98
- Q54L (p.Gln54Leu), NCI-TCGA Cosmic COSV6340, cosmic curated COSV63405, Variant assessed as somatic; moderate impact.
- Q54R (p.Gln54Arg), ExAC rs769793351, gnomAD rs769793351, REVEL 0.19, CADD 21.30
- V55L (p.Val55Leu), rs2524849497, ClinGen CA343228811, ClinVar RCV002787908, REVEL 0.24, CADD 23.00, Uncertain significance, Inborn genetic diseases
- V55E (p.Val55Glu), gnomAD 1-160121238-T-A, REVEL 0.56, CADD 23.30
- V55V (p.Val55Val), rs2101984073, gnomAD 1-160121239-G-A, CADD 10.10
- D56N (p.Asp56Asn), Ensembl rs2101984074
- D56Y (p.Asp56Tyr), gnomAD 1-160121240-G-T, REVEL 0.86, CADD 32.00
- D56D (p.Asp56Asp), rs377335018, gnomAD 1-160121242-C-T, CADD 7.87
- L57P (p.Leu57Pro), rs748802547, ClinGen CA1194106, ClinVar RCV002611592, ExAC rs748802547, REVEL 0.61, CADD 24.20, Uncertain significance, Familial hemiplegic migraine
- L57L (p.Leu57Leu), rs1651388179, gnomAD 1-160121245-G-C, CADD 6.99
- S58T (p.Ser58Thr), rs2524849522, ClinGen CA343228940, ClinVar RCV003587774, Uncertain significance, Familial hemiplegic migraine
- K59T (p.Lys59Thr), rs1367410532, ClinGen CA343228956, ClinVar RCV001049645, TOPMed rs1367410532, REVEL 0.19, CADD 22.40, Uncertain significance, Familial hemiplegic migraine
- K59E (p.Lys59Glu), gnomAD 1-160121249-A-G, REVEL 0.28, CADD 22.40
- G60D (p.Gly60Asp), rs1210388068, ClinGen CA343230242, ClinVar RCV003814016, gnomAD rs1210388068, REVEL 0.95, CADD 33.00, Uncertain significance, Familial hemiplegic migraine
- G60G (p.Gly60Gly), gnomAD 1-160123215-C-A, CADD 13.40
- L61V (p.Leu61Val), gnomAD 1-160123216-C-G, REVEL 0.74, CADD 24.20
- T62I (p.Thr62Ile), Ensembl rs1651474954
- T62S (p.Thr62Ser), rs1651474954, ClinGen CA343230302, ClinVar RCV002979647, AlphaMissense 0.72, MetaLR 0.78, Uncertain significance, Familial hemiplegic migraine
- T62A (p.Thr62Ala), gnomAD 1-160123219-A-G, REVEL 0.55, CADD 23.60
- Q64H (p.Gln64His), rs796052282, ClinGen CA313349, ClinVar RCV000186812, ClinVar RCV000764992, REVEL 0.27, CADD 23.00, Uncertain significance, Inborn genetic diseases; not provided; Migraine, familial hemiplegic, 2
- Q64L (p.Gln64Leu), Ensembl rs1651475147
- Q64K (p.Gln64Lys), gnomAD 1-160123225-C-A, REVEL 0.27, CADD 18.10
- Q64* (p.Gln64Ter), gnomAD 1-160123225-C-T, CADD 36.00
- R65L (p.Arg65Leu), rs187733403, ClinGen CA245145, cosmic curated COSV63404, ClinVar RCV000333542, REVEL 0.60, CADD 22.40, Conflicting interpretations, Developmental and epileptic encephalopathy 98; Inborn genetic diseases; Familial
- R65Q (p.Arg65Gln), rs187733403, ClinGen CA1194140, ClinVar RCV003747494, 1000Genomes rs187733403, REVEL 0.43, CADD 20.90, Uncertain significance, Familial hemiplegic migraine
- R65W (p.Arg65Trp), rs121918619, ClinGen CA256653, cosmic curated COSV63404, ClinVar RCV000013792, REVEL 0.66, CADD 24.40, Uncertain significance, Familial hemiplegic migraine; not provided; Migraine, familial hemiplegic, 2
- R65R (p.Arg65Arg), rs121918619, gnomAD 1-160123228-C-A, CADD 9.38
- Q67E (p.Gln67Glu), gnomAD rs1239361196, REVEL 0.21, CADD 13.40
- D68E (p.Asp68Glu), ExAC rs745431386, TOPMed rs745431386, gnomAD rs745431386, REVEL 0.17, CADD 8.27, Likely benign
- D68N (p.Asp68Asn), rs1651476108, ClinGen CA343230418, ClinVar RCV003586718, AlphaMissense 0.27, MetaLR 0.37, Uncertain significance, Familial hemiplegic migraine
- D68Y (p.Asp68Tyr), rs1651476108, ClinGen CA343230424, ClinVar RCV001205050, ClinVar RCV004768916, AlphaMissense 0.27, MetaLR 0.37, Uncertain significance, not provided; Familial hemiplegic migraine
- D68D (p.Asp68Asp), rs745431386, gnomAD 1-160123239-C-T, CADD 6.08
Public ATP1A2 analysis runs
- ATP1A2 analysis run — ATP1A2 (1,218 variants) — completed 2026-08-18