AQP2 (Aquaporin-2) variants and mutations
AQP2 (also known as Aquaporin-2) is a human protein-coding gene encoding an aquaporin-2 protein. It is inserted into the collecting-duct apical membrane in response to vasopressin, allowing water reabsorption and concentration of urine. Pathogenic variants cause nephrogenic diabetes insipidus, usually recessive for loss-of-function alleles and sometimes dominant through abnormal intracellular trafficking. This analysis covers 675 AQP2 variants and mutations. Of these, 89% have computational variant effect predictions. Disease context includes diabetes insipidus, nephrogenic, autosomal, nephrogenic diabetes insipidus, and neurodegenerative disease. Example AQP2 variants include M1I, W2*, and W2S.
Variant analysis overview
- Gene: AQP2
- Protein: Aquaporin-2
- UniProt accession: P41181
- Organism: Homo sapiens
- Variants analyzed: 675
- Variant scope: all variants
- Completed: 2026-08-19
Variant and mutation evidence
- Variant composition: 337 unspecified-consequence records; 184 missense variants; 123 synonymous variants; 19 frameshift variants; 1 in-frame deletions; 3 splice-region variants; 6 stop-gained variants; 2 substitution
- Prediction scores: 601 variants have prediction scores (89% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: diabetes insipidus, nephrogenic, autosomal, nephrogenic diabetes insipidus, neurodegenerative disease, diabetes insipidus, dermatophytosis, allergic rhinitis, fungal infectious disease, epilepsy, tinea pedis, Epidermal thickening, hereditary disease, alcohol drinking.
Protein structure and variant hotspots
- Protein features: 6 transmembrane segments; 2 post-translational modification sites.
- Structural context: 321 variants have structural context.
- PTM context: 3 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, MaveDB, LitVar.
Notable AQP2 variants
Examples include M1I, W2*, W2S, E3*, E3K, E3Q, E3E, L4P. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1I (p.Met1Ile), rs1288385043, ClinGen CA384771345, ClinVar RCV001293732, MetaLR 0.52, MetaSVM 0.04, Pathogenic, Nephrogenic diabetes insipidus
- W2* (p.Trp2Ter), TOPMed rs1382799709, gnomAD rs1382799709, CADD 38.00
- W2S (p.Trp2Ser), TOPMed rs1382799709, gnomAD rs1382799709, REVEL 0.65, CADD 25.00
- E3* (p.Glu3Ter), NCI-TCGA Cosmic COSV5222, Variant assessed as somatic; high impact.
- E3K (p.Glu3Lys), rs779279677, NCI-TCGA Cosmic COSV5222, ExAC rs779279677, gnomAD rs779279677, REVEL 0.79, CADD 29.10, Uncertain significance, Diabetes insipidus, nephrogenic, autosomal
- E3Q (p.Glu3Gln), gnomAD 12-49950837-G-C, REVEL 0.76, CADD 26.90
- E3E (p.Glu3Glu), rs748337255, gnomAD 12-49950839-G-A, CADD 8.58
- L4P (p.Leu4Pro), ESP rs372883230, TOPMed rs372883230, gnomAD rs372883230, REVEL 0.84, CADD 28.20
- L4V (p.Leu4Val), TOPMed rs1365398150, gnomAD rs1365398150, REVEL 0.20, CADD 18.40, Uncertain significance, not provided
- R5C (p.Arg5Cys), rs772585705, ClinGen CA6559124, NCI-TCGA Cosmic COSV5223, ClinVar RCV002598813, REVEL 0.41, CADD 22.80, Uncertain significance, not provided; Diabetes insipidus, nephrogenic, autosomal
- R5H (p.Arg5His), rs148006652, ClinGen CA6559125, ClinVar RCV002647707, ClinVar RCV002663947, REVEL 0.61, CADD 24.70, Uncertain significance, Inborn genetic diseases; not provided
- R5R (p.Arg5Arg), rs761283952, gnomAD 12-49950845-C-A, CADD 5.99
- S6P (p.Ser6Pro), gnomAD 12-49950846-T-C, REVEL 0.78, CADD 26.90
- S6F (p.Ser6Phe), gnomAD 12-49950847-C-T, REVEL 0.83, CADD 25.80
- I7T (p.Ile7Thr), rs1592814511, ClinGen CA384771415, ClinVar RCV003121408, Ensembl rs1592814511, REVEL 0.30, CADD 20.50, Uncertain significance, not provided
- I7V (p.Ile7Val), TOPMed rs1278004193, gnomAD rs1278004193, REVEL 0.19, CADD 9.43
- A8D (p.Ala8Asp), TOPMed rs1237811033, gnomAD rs1237811033, REVEL 0.53, CADD 25.30
- A8T (p.Ala8Thr), TOPMed rs1354001307, gnomAD rs1354001307, REVEL 0.34, CADD 22.60
- A8S (p.Ala8Ser), gnomAD 12-49950852-G-T, REVEL 0.27, CADD 21.30
- A8P (p.Ala8Pro), gnomAD 12-49950852-G-C, REVEL 0.35, CADD 22.50
- A8A (p.Ala8Ala), rs1592814524, gnomAD 12-49950854-C-T, CADD 10.40
- F9L (p.Phe9Leu), NCI-TCGA Cosmic COSV9955, Variant assessed as somatic; moderate impact.
- F9S (p.Phe9Ser), Ensembl rs1224587357
- F9F (p.Phe9Phe), rs187754589, gnomAD 12-49950857-C-T, CADD 10.50
- S10F (p.Ser10Phe), gnomAD 12-49950859-C-T, REVEL 0.38, CADD 19.10
- S10S (p.Ser10Ser), rs777139117, gnomAD 12-49950860-C-T, CADD 11.70
- R11K (p.Arg11Lys), rs148085137, ClinGen CA6559129, ClinVar RCV001111885, 1000Genomes rs148085137, REVEL 0.48, CADD 22.20, Uncertain significance, Diabetes insipidus, nephrogenic, autosomal
- R11R (p.Arg11Arg), rs1394641835, gnomAD 12-49950863-G-A, CADD 9.87
- A12T (p.Ala12Thr), Ensembl rs1947323187, REVEL 0.77, CADD 27.50
- A12S (p.Ala12Ser), gnomAD 12-49950864-G-T, REVEL 0.73, CADD 26.20
- A12A (p.Ala12Ala), gnomAD 12-49950866-T-G, CADD 1.00
- V13V (p.Val13Val), rs61733029, gnomAD 12-49950869-G-A, CADD 9.28
- F14L (p.Phe14Leu), ExAC rs775148085, TOPMed rs775148085, gnomAD rs775148085, REVEL 0.21, CADD 0.67, Likely benign
- F14I (p.Phe14Ile), gnomAD 12-49950870-T-A, REVEL 0.23, CADD 16.50
- F14F (p.Phe14Phe), rs775148085, gnomAD 12-49950872-C-T, CADD 2.61
- A15T (p.Ala15Thr), ExAC rs762574510, TOPMed rs762574510, gnomAD rs762574510, REVEL 0.43, CADD 18.90, Uncertain significance, not provided; Diabetes insipidus, nephrogenic, autosomal
- A15S (p.Ala15Ser), gnomAD 12-49950873-G-T, REVEL 0.45, CADD 17.20
- E16G (p.Glu16Gly), gnomAD 12-49950877-A-G, REVEL 0.92, CADD 29.70
- F17L (p.Phe17Leu), ExAC rs763919973, gnomAD rs763919973, NCI-TCGA Cosmic COSV5222, REVEL 0.71, CADD 23.10, Variant assessed as somatic; moderate impact.
- L18R (p.Leu18Arg), TOPMed rs1592814548, REVEL 0.89, CADD 27.20
- A19T (p.Ala19Thr), ExAC rs751311089, gnomAD rs751311089
- A19V (p.Ala19Val), TOPMed rs1349575785
- A19S (p.Ala19Ser), gnomAD 12-49950885-G-T, REVEL 0.60, CADD 24.30
- T20I (p.Thr20Ile), TOPMed rs1323425355, gnomAD rs1323425355, REVEL 0.93, CADD 25.10, Uncertain significance, Inborn genetic diseases
- T20A (p.Thr20Ala), gnomAD 12-49950888-A-G, REVEL 0.89, CADD 25.90
- T20T (p.Thr20Thr), gnomAD 12-49950890-A-T, CADD 0.97
- L21F (p.Leu21Phe), ExAC rs757280714, TOPMed rs757280714, gnomAD rs757280714, REVEL 0.24, CADD 18.80, Uncertain significance, not provided
- L21P (p.Leu21Pro), rs1393300849, ClinGen CA384771580, ClinVar RCV000722991, TOPMed rs1393300849, REVEL 0.76, CADD 24.40, Uncertain significance, not provided
- L21V (p.Leu21Val), ExAC rs757280714, TOPMed rs757280714, gnomAD rs757280714, REVEL 0.43, CADD 18.20
- L21H (p.Leu21His), rs1947323487, gnomAD 12-49950886-C-CCA, CADD 25.70
- L21L (p.Leu21Leu), rs147136099, gnomAD 12-49950893-C-G, CADD 8.95
- L22V (p.Leu22Val), rs104894336, ClinGen CA127482, ClinVar RCV000019416, ClinVar RCV006461183, REVEL 0.49, CADD 12.80, Uncertain significance, not provided; Diabetes insipidus, nephrogenic, autosomal
- L22P (p.Leu22Pro), gnomAD 12-49950894-CT-C, CADD 26.50
- L22L (p.Leu22Leu), gnomAD 12-49950896-C-G, CADD 9.48
- F23L (p.Phe23Leu), NCI-TCGA Cosmic COSV9955, gnomAD rs1947323649, REVEL 0.65, CADD 27.60, Variant assessed as somatic; moderate impact.
- F23F (p.Phe23Phe), rs779085450, gnomAD 12-49950899-C-T, CADD 0.50
- V24I (p.Val24Ile), rs200706192, ClinGen CA6559139, ClinVar RCV000375579, ClinVar RCV000933479, REVEL 0.55, CADD 23.20, Conflicting interpretations, not provided; Diabetes insipidus, nephrogenic, autosomal
- V24V (p.Val24Val), gnomAD 12-49950902-C-G, CADD 9.71
- F26F (p.Phe26Phe), rs758661503, gnomAD 12-49950908-T-C, CADD 7.03
- G27R (p.Gly27Arg), ExAC rs778267384, gnomAD rs778267384, REVEL 0.93, CADD 28.30
- L28F (p.Leu28Phe), gnomAD rs1333138865, REVEL 0.54, CADD 24.10, Uncertain significance, in NDI2
- L28H (p.Leu28His), TOPMed rs1947323748
- L28I (p.Leu28Ile), gnomAD rs1333138865, REVEL 0.33, CADD 19.40, Uncertain significance, not provided; Diabetes insipidus, nephrogenic, autosomal
- L28P (p.Leu28Pro), UniProt VAR 015240, Pathogenic, in NDI2
- L28V (p.Leu28Val), gnomAD rs1333138865, Uncertain significance, in NDI2
- L28L (p.Leu28Leu), rs373926562, gnomAD 12-49950914-C-T, CADD 0.42
- G29S (p.Gly29Ser), rs964170650, ClinGen CA236731096, ClinVar RCV002947905, ClinVar RCV003235748, REVEL 0.86, CADD 27.00, Conflicting interpretations, Nephrogenic diabetes insipidus; not provided; Diabetes insipidus, nephrogenic, a
- G29V (p.Gly29Val), gnomAD 12-49950916-G-T, REVEL 0.93, CADD 26.90
- G29G (p.Gly29Gly), gnomAD 12-49950917-C-T, CADD 10.60
- S30P (p.Ser30Pro), gnomAD 12-49950918-T-C, REVEL 0.85, CADD 26.50
- S30C (p.Ser30Cys), gnomAD 12-49950919-C-G, REVEL 0.80, CADD 25.50
- A31G (p.Ala31Gly), TOPMed rs1304396038, gnomAD rs1304396038, REVEL 0.74, CADD 24.90
- A31T (p.Ala31Thr), Ensembl rs1947323866, Uncertain significance, Nephrogenic diabetes insipidus
- A31V (p.Ala31Val), gnomAD 12-49950922-C-T, REVEL 0.65, CADD 22.50
- A31A (p.Ala31Ala), rs771261931, gnomAD 12-49950923-C-T, CADD 9.75
- L32I (p.Leu32Ile), TOPMed rs1947323940, Uncertain significance, Diabetes insipidus, nephrogenic, autosomal
- N33I (p.Asn33Ile), Ensembl rs2137144210
- N33C (p.Asn33Cys), rs772201159, gnomAD 12-49950918-TCTGC, CADD 28.60
- N33S (p.Asn33Ser), gnomAD 12-49950928-A-G, REVEL 0.21, CADD 16.20
- N33N (p.Asn33Asn), gnomAD 12-49950929-C-T, CADD 8.44
- W34* (p.Trp34Ter), ExAC rs777037742, gnomAD rs777037742, CADD 38.00
- W34R (p.Trp34Arg), gnomAD 12-49950930-T-C, REVEL 0.75, CADD 27.70
- W34C (p.Trp34Cys), gnomAD 12-49950932-G-T, REVEL 0.76, CADD 29.80
- P35S (p.Pro35Ser), ExAC rs746338782, gnomAD rs746338782, REVEL 0.41, CADD 17.90
- P35T (p.Pro35Thr), ExAC rs746338782, gnomAD rs746338782
- P35A (p.Pro35Ala), gnomAD 12-49950933-C-G, REVEL 0.26, CADD 16.60
- Q36* (p.Gln36Ter), rs1947324005, ClinGen CA384771758, ClinVar RCV001900674, TOPMed rs1947324005, CADD 33.00, Pathogenic
- Q36R (p.Gln36Arg), Ensembl rs1947324028, REVEL 0.16, CADD 6.45
- A37S (p.Ala37Ser), Ensembl rs1947324056
- A37V (p.Ala37Val), TOPMed rs1947324078, gnomAD rs1947324078, REVEL 0.05, CADD 14.00, Uncertain significance, Nephrogenic diabetes insipidus
- L38C (p.Leu38Cys), gnomAD 12-49950939-GC-G, CADD 16.10
- L38V (p.Leu38Val), gnomAD 12-49950942-C-G, REVEL 0.04, CADD 8.19
- L38L (p.Leu38Leu), rs774952238, gnomAD 12-49950944-G-A, CADD 7.38
- P39H (p.Pro39His), Ensembl rs1947324124, REVEL 0.39, CADD 24.80
- P39S (p.Pro39Ser), gnomAD 12-49950945-C-T, REVEL 0.35, CADD 22.50
- S40C (p.Ser40Cys), rs2547996975, ClinGen CA384771807, ClinVar RCV004420030, Uncertain significance, Inborn genetic diseases
- V41L (p.Val41Leu), TOPMed rs1947324146
- V41V (p.Val41Val), gnomAD 12-49950953-G-A, CADD 6.12
- L42P (p.Leu42Pro), 1000Genomes rs762664471, ExAC rs762664471, gnomAD rs762664471, REVEL 0.77, CADD 27.00
- L42V (p.Leu42Val), TOPMed rs1947324164
- L42L (p.Leu42Leu), rs1240491953, gnomAD 12-49950956-A-G, CADD 8.75
- Q43* (p.Gln43Ter), rs1481158831, ClinGen CA384771830, ClinVar RCV001939528, ClinVar RCV002507699, CADD 37.00, Pathogenic
- Q43P (p.Gln43Pro), ExAC rs763727714, gnomAD rs763727714, REVEL 0.86, CADD 25.80
- Q43R (p.Gln43Arg), ExAC rs763727714, gnomAD rs763727714, REVEL 0.73, CADD 25.40
- Q43D (p.Gln43Asp), rs1337669269, gnomAD 12-49950955-TAC-T, CADD 25.90
- Q43E (p.Gln43Glu), gnomAD 12-49950957-C-G, REVEL 0.71, CADD 24.30
- I44T (p.Ile44Thr), rs1248655050, ClinGen CA384771960, ClinVar RCV004420031, TOPMed rs1248655050, REVEL 0.76, CADD 23.60, Uncertain significance, Inborn genetic diseases
- A45G (p.Ala45Gly), TOPMed rs1284823222, gnomAD rs1284823222, REVEL 0.74, CADD 22.10
- A45T (p.Ala45Thr), NCI-TCGA Cosmic COSV5223, Ensembl rs1947324308, REVEL 0.76, CADD 23.30, Variant assessed as somatic; moderate impact.
- M46I (p.Met46Ile), ExAC rs767301067, gnomAD rs767301067, REVEL 0.26, CADD 14.20
- M46L (p.Met46Leu), ExAC rs761515066, gnomAD rs761515066, REVEL 0.12, AlphaMissense 0.17
- A47E (p.Ala47Glu), TOPMed rs995684800, gnomAD rs995684800, REVEL 0.77, AlphaMissense 0.22, Likely pathogenic, in NDI2
- A47V (p.Ala47Val), rs995684800, ClinGen CA236731189, NCI-TCGA Cosmic COSV5223, ClinVar RCV003558579, REVEL 0.77, CADD 23.90, Likely pathogenic, not provided; Nephrogenic diabetes insipidus
- A47A (p.Ala47Ala), gnomAD 12-49950971-G-T, AlphaMissense 0.12, MetaLR 0.85
- F48I (p.Phe48Ile), gnomAD rs1172724582, REVEL 0.80, CADD 24.30
- G49del (p.Gly49del), rs1354952791, gnomAD 12-49950973-TTGG-, CADD 16.80
- G49D (p.Gly49Asp), gnomAD 12-49950976-G-A, REVEL 0.89, CADD 24.50
- L50L (p.Leu50Leu), rs756096963, gnomAD 12-49950980-G-A, CADD 3.08
- G51C (p.Gly51Cys), NCI-TCGA Cosmic COSV5223, REVEL 0.55, CADD 24.10, Variant assessed as somatic; moderate impact.
- G51S (p.Gly51Ser), gnomAD 12-49950981-G-A, REVEL 0.21, CADD 22.40
- G51V (p.Gly51Val), gnomAD 12-49950982-G-T, REVEL 0.24, CADD 16.00
- G51G (p.Gly51Gly), rs1592814622, gnomAD 12-49950983-T-G, CADD 0.45
- I52T (p.Ile52Thr), rs2137144293, ClinGen CA384772013, ClinVar RCV001580625, Ensembl rs2137144293, REVEL 0.62, CADD 22.00, Uncertain significance, Diabetes insipidus, nephrogenic, autosomal
- G53C (p.Gly53Cys), TOPMed rs1947324535, Uncertain significance, Diabetes insipidus, nephrogenic, autosomal
- G53G (p.Gly53Gly), gnomAD 12-49950989-C-A, AlphaMissense 0.09, MetaLR 0.74
- T54I (p.Thr54Ile), TOPMed rs1466275664, gnomAD rs1466275664, REVEL 0.81, CADD 24.00
- T54N (p.Thr54Asn), TOPMed rs1466275664, gnomAD rs1466275664
- T54P (p.Thr54Pro), Ensembl rs1592814625
- T54T (p.Thr54Thr), rs143497314, gnomAD 12-49950992-C-T, CADD 6.96
- L55L (p.Leu55Leu), rs752819840, gnomAD 12-49950993-C-T, CADD 5.95
- L55P (p.Leu55Pro), gnomAD 12-49950994-T-C, REVEL 0.92, CADD 26.70
- V56I (p.Val56Ile), gnomAD rs1396199369, REVEL 0.37, CADD 23.00
- V56V (p.Val56Val), rs982837638, gnomAD 12-49950998-A-G, AlphaMissense 0.06, MetaLR 0.77
- Q57P (p.Gln57Pro), rs28931580, ClinGen CA127486, ClinVar RCV000019420, ClinVar RCV001039718, REVEL 0.90, CADD 25.20, Pathogenic/Likely pathogenic, not provided; Nephrogenic diabetes insipidus; Diabetes insipidus, nephrogenic, a
- A58G (p.Ala58Gly), ExAC rs575346865, TOPMed rs575346865, gnomAD rs575346865, REVEL 0.39, CADD 15.20, Uncertain significance, Inborn genetic diseases
- A58T (p.Ala58Thr), ESP rs145685755, ExAC rs145685755, TOPMed rs145685755, gnomAD rs145685755, REVEL 0.12, CADD 3.88
- A58V (p.Ala58Val), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- A58D (p.Ala58Asp), gnomAD 12-49951003-C-A, REVEL 0.64, CADD 22.90
- L59L (p.Leu59Leu), gnomAD 12-49951005-C-T, AlphaMissense 0.06, MetaLR 0.80
- G60S (p.Gly60Ser), rs1014984131, NCI-TCGA Cosmic COSV5222, Ensembl rs1014984131, AlphaMissense 0.45, MetaLR 0.91, Variant assessed as somatic; moderate impact.
- G60D (p.Gly60Asp), gnomAD 12-49951009-G-A, REVEL 0.94, CADD 24.60
- G60A (p.Gly60Ala), gnomAD 12-49951009-G-C, REVEL 0.89, AlphaMissense 0.14
- G60G (p.Gly60Gly), rs370848842, gnomAD 12-49951010-C-T, CADD 5.72
- I62K (p.Ile62Lys), TOPMed rs1308492971, gnomAD rs1308492971, REVEL 0.71, CADD 22.80
- I62L (p.Ile62Leu), ExAC rs781600142, gnomAD rs781600142, REVEL 0.44, CADD 0.25
- I62T (p.Ile62Thr), TOPMed rs1308492971, gnomAD rs1308492971, REVEL 0.52, CADD 19.60
- I62V (p.Ile62Val), gnomAD 12-49951014-A-G, REVEL 0.19, CADD 0.00
- S63N (p.Ser63Asn), ExAC rs746416707, TOPMed rs746416707, gnomAD rs746416707, REVEL 0.71, CADD 24.30
- S63R (p.Ser63Arg), 1000Genomes rs200279968, ExAC rs200279968, TOPMed rs200279968, gnomAD rs200279968, REVEL 0.69, CADD 8.74, Likely benign
- S63C (p.Ser63Cys), gnomAD 12-49951017-A-T, REVEL 0.89, AlphaMissense 0.14
- S63S (p.Ser63Ser), rs200279968, gnomAD 12-49951019-C-T, CADD 0.47
- G64R (p.Gly64Arg), rs104894326, ClinGen CA127468, NCI-TCGA Cosmic COSV5222, ClinVar RCV000518067, REVEL 0.95, CADD 25.30, Pathogenic/Likely pathogenic, not provided; Nephrogenic diabetes insipidus; Diabetes insipidus, nephrogenic, a
- G64V (p.Gly64Val), gnomAD 12-49951021-G-T, REVEL 0.94, CADD 24.80
- A65P (p.Ala65Pro), 1000Genomes rs544999593, ExAC rs544999593, gnomAD rs544999593, REVEL 0.86, CADD 25.10
- A65T (p.Ala65Thr), 1000Genomes rs544999593, ExAC rs544999593, gnomAD rs544999593, REVEL 0.72, CADD 25.20
- A65V (p.Ala65Val), TOPMed rs147174725, gnomAD rs147174725, REVEL 0.81, CADD 24.40
- H66Y (p.His66Tyr), gnomAD rs1256982565, REVEL 0.94, CADD 24.00
- H66D (p.His66Asp), gnomAD 12-49951026-C-G, REVEL 0.94, CADD 24.60
- I67T (p.Ile67Thr), ExAC rs773903320, REVEL 0.89, CADD 24.90
- N68S (p.Asn68Ser), rs104894331, ClinGen CA127474, ClinVar RCV000019412, UniProt VAR 015242, AlphaMissense 0.96, MetaLR 0.98, Pathogenic, Diabetes insipidus, nephrogenic, autosomal
- N68T (p.Asn68Thr), ExAC rs104894331, gnomAD rs104894331, REVEL 0.91, AlphaMissense 0.96, Pathogenic, in NDI2
- N68N (p.Asn68Asn), rs57915981, gnomAD 12-49951034-C-T, AlphaMissense 0.10, MetaLR 0.82
- N68K (p.Asn68Lys), gnomAD 12-49951034-C-A, REVEL 0.75, CADD 19.40
- P69L (p.Pro69Leu), gnomAD 12-49951036-C-T, REVEL 0.95, CADD 24.30
- P69P (p.Pro69Pro), gnomAD 12-49951037-T-A, CADD 0.14
- A70D (p.Ala70Asp), UniProt VAR 062585, Pathogenic, in NDI2
- A70V (p.Ala70Val), NCI-TCGA Cosmic COSV5223, Variant assessed as somatic; moderate impact., in NDI2
- A70A (p.Ala70Ala), rs139893949, gnomAD 12-49951040-C-A, CADD 1.07
- V71A (p.Val71Ala), TOPMed rs1947325185
- V71L (p.Val71Leu), TOPMed rs149659001, gnomAD rs149659001, REVEL 0.87, CADD 26.10, Pathogenic, in NDI2
- V71M (p.Val71Met), rs149659001, ClinGen CA236731400, ClinVar RCV000516325, ClinVar RCV001329304, REVEL 0.87, CADD 27.20, Pathogenic/Likely pathogenic, not provided; Diabetes insipidus, nephrogenic, autosomal
- V71V (p.Val71Val), gnomAD 12-49951043-G-T, CADD 10.30
- V73G (p.Val73Gly), rs1451418775, gnomAD 12-49951045-CTG-C, CADD 25.60
- V73V (p.Val73Val), gnomAD 12-49951049-G-A, CADD 9.26
- A74T (p.Ala74Thr), gnomAD 12-49951050-G-A, REVEL 0.85, CADD 29.10
- A74A (p.Ala74Ala), gnomAD 12-49951052-C-T, CADD 10.70
- C75F (p.Cys75Phe), NCI-TCGA Cosmic COSV5223, Variant assessed as somatic; moderate impact.
- C75G (p.Cys75Gly), rs193922494, ClinGen CA260118, ClinVar RCV000029341, Ensembl rs193922494, AlphaMissense 0.47, MetaLR 0.68, Likely pathogenic, Nephrogenic diabetes insipidus
- C75S (p.Cys75Ser), TOPMed rs144443773, gnomAD rs144443773
- C75Y (p.Cys75Tyr), TOPMed rs144443773, gnomAD rs144443773, REVEL 0.10, CADD 20.20
Public AQP2 analysis runs
- AQP2 analysis run — AQP2 (675 variants) — completed 2026-08-19