ANKRD1 (Q15327) variants and mutations
ANKRD1 (also known as Q15327) is a human protein-coding gene encoding an ankyrin repeat domain-containing protein 1 protein. It localizes to the cardiac sarcomere and nucleus, where it participates in mechanosensing and stress-responsive transcription. Rare pathogenic variants have been associated with dilated and hypertrophic cardiomyopathy, although penetrance and variant-specific evidence can vary. This analysis covers 605 ANKRD1 variants and mutations. Of these, 80% have computational variant effect predictions. Disease context includes familial isolated dilated cardiomyopathy, alcohol drinking, and tooth disorder. Example ANKRD1 variants include M1I, M1V, and M2T.
Variant analysis overview
- Gene: ANKRD1
- Protein: Q15327
- UniProt accession: Q15327
- Organism: Homo sapiens
- Variants analyzed: 605
- Variant scope: all variants
- Completed: 2026-08-21
Variant and mutation evidence
- Variant composition: 459 unspecified-consequence records; 69 synonymous variants; 57 missense variants; 3 in-frame deletions; 9 frameshift variants; 4 stop-gained variants; 3 splice-region variants; 1 substitution
- Prediction scores: 484 variants have prediction scores (80% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: familial isolated dilated cardiomyopathy, alcohol drinking, tooth disorder, schizophrenia, dilated cardiomyopathy, ankrd1-related dilated cardiomyopathy, Abnormality of the cardiovascular system, refractive error, autosomal dominant dilated cardiomyopathy, cardiomyopathy, familial hypertrophic cardiomyopathy, Rare familial disorder with hypertrophic cardiomyopathy.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable ANKRD1 variants
Examples include M1I, M1V, M2T, V3A, K5Q, E7D, E8K, V10F. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1I (p.Met1Ile), rs188706671, ClinGen CA377554435, ClinVar RCV001700568, ClinGen CA5598881, MetaLR 0.20, MetaSVM -0.66, Uncertain significance, not provided
- M1V (p.Met1Val), rs772918277, ClinGen CA5598884, ClinVar RCV001917693, MetaLR 0.24, MetaSVM -0.56, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- M2T (p.Met2Thr), ExAC rs768122383, gnomAD rs768122383, REVEL 0.21, CADD 22.80, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- V3A (p.Val3Ala), rs2492964562, ClinGen CA377554406, ClinVar RCV002301783, NCI-TCGA TCGA novel, REVEL 0.14, CADD 23.20, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- K5Q (p.Lys5Gln), rs2492964545, ClinGen CA377554393, ClinVar RCV003046846, REVEL 0.04, CADD 18.20, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- E7D (p.Glu7Asp), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
- E8K (p.Glu8Lys), rs1847431695, ClinGen CA377554354, ClinVar RCV002446305, gnomAD rs1847431695, REVEL 0.20, CADD 23.40, Uncertain significance, Cardiovascular phenotype
- V10F (p.Val10Phe), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- V10I (p.Val10Ile), rs757040674, ClinGen CA5598856, ClinVar RCV003071722, ClinVar RCV003443117, REVEL 0.35, CADD 27.20, Uncertain significance, not provided; Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- K14N (p.Lys14Asn), NCI-TCGA Cosmic COSV6331, REVEL 0.20, CADD 24.10, Variant assessed as somatic; moderate impact.
- N15H (p.Asn15His), 1000Genomes rs571287478, ExAC rs571287478, TOPMed rs571287478, gnomAD rs571287478, REVEL 0.10, CADD 18.60
- G16C (p.Gly16Cys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- G16V (p.Gly16Val), TOPMed rs1847422812, Uncertain significance, Cardiovascular phenotype
- N17D (p.Asn17Asp), rs1057522674, ClinGen CA16605734, ClinVar RCV000424331, ClinVar RCV001313194, REVEL 0.07, CADD 9.40, Uncertain significance, not provided; ANKRD1-related dilated cardiomyopathy
- G18A (p.Gly18Ala), rs756262750, ClinGen CA5598852, ClinVar RCV002347259, ClinVar RCV006470831, REVEL 0.04, CADD 7.30, Uncertain significance, Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- G18R (p.Gly18Arg), ExAC rs778081649, gnomAD rs778081649, REVEL 0.07, CADD 15.10
- G18W (p.Gly18Trp), ExAC rs778081649, gnomAD rs778081649
- E19D (p.Glu19Asp), rs1431425358, ClinGen CA377554121, ClinVar RCV001772856, ClinVar RCV003642973, REVEL 0.06, CADD 0.07, Conflicting interpretations, Cardiovascular phenotype; not provided; ANKRD1-related dilated cardiomyopathy
- E19K (p.Glu19Lys), rs886047480, ClinGen CA377554130, ClinVar RCV001306664, TOPMed rs886047480, REVEL 0.06, CADD 18.70, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- E19Q (p.Glu19Gln), rs886047480, ClinGen CA10632855, ClinVar RCV000372006, ClinVar RCV005659890, REVEL 0.07, CADD 16.90, Uncertain significance, Primary dilated cardiomyopathy; Cardiovascular phenotype
- A20E (p.Ala20Glu), rs775935256, ClinGen CA5598851, ClinVar RCV003090215, ExAC rs775935256, REVEL 0.08, CADD 14.60, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- A20V (p.Ala20Val), ExAC rs775935256, TOPMed rs775935256, gnomAD rs775935256, REVEL 0.09, CADD 16.30, Likely benign, Cardiovascular phenotype
- G21E (p.Gly21Glu), NCI-TCGA TCGA novel, Ensembl rs1847422439, REVEL 0.29, CADD 18.30, Variant assessed as somatic; moderate impact.
- E22K (p.Glu22Lys), rs1589510880, ClinGen CA377554096, ClinVar RCV000811314, Ensembl rs1589510880, REVEL 0.10, CADD 22.20, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- P25H (p.Pro25His), rs1191329876, ClinGen CA377554048, ClinVar RCV003171194, ClinVar RCV006473810, REVEL 0.23, CADD 24.50, Uncertain significance, Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- P25L (p.Pro25Leu), gnomAD rs1191329876, REVEL 0.29, CADD 23.40, Uncertain significance
- P25S (p.Pro25Ser), ExAC rs752073000, gnomAD rs752073000, REVEL 0.24, CADD 22.30
- E26D (p.Glu26Asp), Ensembl rs1589510867
- E26G (p.Glu26Gly), Ensembl rs1589510870
- D27E (p.Asp27Glu), Ensembl rs1589510864
- D27Y (p.Asp27Tyr), rs1847422222, ClinGen CA377554025, ClinVar RCV001760763, Ensembl rs1847422222, AlphaMissense 0.18, MetaLR 0.31, Uncertain significance, not provided
- R29G (p.Arg29Gly), ExAC rs766683591, gnomAD rs766683591, REVEL 0.14, CADD 22.90
- D30N (p.Asp30Asn), gnomAD rs1589510859, REVEL 0.08, CADD 17.70, Uncertain significance
- D30Y (p.Asp30Tyr), rs1589510859, ClinGen CA377553981, ClinVar RCV002376061, gnomAD rs1589510859, REVEL 0.12, CADD 22.90, Uncertain significance, Cardiovascular phenotype
- G31A (p.Gly31Ala), ExAC rs763320656, TOPMed rs763320656, gnomAD rs763320656, Uncertain significance
- G31E (p.Gly31Glu), rs763320656, ClinGen CA5598846, ClinVar RCV000422635, ClinVar RCV002374656, REVEL 0.37, CADD 27.00, Uncertain significance, Cardiovascular phenotype; not provided
- E32D (p.Glu32Asp), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
- E32Q (p.Glu32Gln), TOPMed rs1417348160, gnomAD rs1417348160, REVEL 0.06, CADD 16.90, Uncertain significance, Cardiovascular phenotype
- Y33* (p.Tyr33Ter), rs2492962826, ClinGen CA377553932, ClinVar RCV002383121, Uncertain significance
- Y33C (p.Tyr33Cys), rs1460361884, ClinGen CA377553940, ClinVar RCV003644224, gnomAD rs1460361884, REVEL 0.61, CADD 31.00, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- Y33H (p.Tyr33His), rs1847421976, ClinGen CA377553943, ClinVar RCV001047453, ClinVar RCV005660021, AlphaMissense 0.91, MetaLR 0.44, Uncertain significance, Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- E34* (p.Glu34Ter), rs1130407, NCI-TCGA Cosmic COSV1007, Ensembl rs1130407, CADD 38.00, Variant assessed as somatic; high impact.
- A35G (p.Ala35Gly), 1000Genomes rs551198213, ExAC rs551198213, gnomAD rs551198213, REVEL 0.22, CADD 23.40
- A35V (p.Ala35Val), 1000Genomes rs551198213, ExAC rs551198213, gnomAD rs551198213, REVEL 0.22, CADD 24.70
- A36T (p.Ala36Thr), TOPMed rs1157286519, gnomAD rs1157286519, REVEL 0.20, CADD 22.70
- A36V (p.Ala36Val), ExAC rs771582860, gnomAD rs771582860, REVEL 0.24, CADD 24.40
- V37A (p.Val37Ala), ExAC rs774292804, TOPMed rs774292804, gnomAD rs774292804, REVEL 0.38, CADD 22.90
- V37I (p.Val37Ile), rs1401851050, ClinGen CA377553891, ClinVar RCV001256725, ClinVar RCV003528282, REVEL 0.08, CADD 17.30, Uncertain significance, ANKRD1-related dilated cardiomyopathy; Hypertrophic cardiomyopathy 1
- T38I (p.Thr38Ile), rs770642356, ClinGen CA5598837, ClinVar RCV003870801, ExAC rs770642356, REVEL 0.09, CADD 22.30, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- L39S (p.Leu39Ser), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
- L39V (p.Leu39Val), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
- E40K (p.Glu40Lys), rs1316020181, ClinGen CA377553852, ClinVar RCV001767407, ClinVar RCV006557663, AlphaMissense 0.59, MetaLR 0.30, Uncertain significance, not provided; ANKRD1-related dilated cardiomyopathy
- E40Q (p.Glu40Gln), rs1316020181, ClinGen CA377553856, ClinVar RCV001327312, TOPMed rs1316020181, REVEL 0.32, AlphaMissense 0.59, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- K41R (p.Lys41Arg), rs1181229749, ClinGen CA377553830, ClinVar RCV001921834, gnomAD rs1181229749, AlphaMissense 0.14, MetaLR 0.40, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- Q42R (p.Gln42Arg), rs1408164414, ClinGen CA377553804, ClinVar RCV001765165, ClinVar RCV002425042, REVEL 0.07, CADD 22.70, Uncertain significance, not provided; Cardiovascular phenotype
- D44E (p.Asp44Glu), rs375587589, ESP rs375587589, ExAC rs375587589, TOPMed rs375587589, REVEL 0.38, CADD 22.60, Uncertain significance, not provided; Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- D44G (p.Asp44Gly), rs749040843, ClinGen CA5598836, ClinVar RCV000413576, ClinVar RCV001836810, REVEL 0.27, CADD 23.80, Uncertain significance, Cardiovascular phenotype; not specified; not provided
- L45Q (p.Leu45Gln), ExAC rs748357650
- L45V (p.Leu45Val), rs372030578, ClinGen CA5598834, ClinVar RCV000852626, ClinVar RCV001811508, REVEL 0.08, CADD 20.40, Conflicting interpretations, not provided; ANKRD1-related dilated cardiomyopathy; Cardiovascular phenotype
- K46M (p.Lys46Met), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- T47A (p.Thr47Ala), TOPMed rs1847421185, REVEL 0.06, CADD 23.30
- T47I (p.Thr47Ile), rs727502891, ClinGen CA175253, ClinVar RCV000150161, ClinVar RCV001326574, REVEL 0.19, CADD 27.10, Uncertain significance, not specified; ANKRD1-related dilated cardiomyopathy
- L48P (p.Leu48Pro), Ensembl rs1564574999
- L48V (p.Leu48Val), rs2492962665, ClinGen CA377553667, ClinVar RCV002392023, Uncertain significance, Cardiovascular phenotype
- L49P (p.Leu49Pro), ESP rs145358212, TOPMed rs145358212, REVEL 0.10, CADD 19.20, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- A50D (p.Ala50Asp), rs2492962643, ClinGen CA377553633, ClinVar RCV003644072, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- A50P (p.Ala50Pro), rs28730751, ClinGen CA136820, ClinVar RCV000038843, ClinVar RCV000250806, REVEL 0.06, AlphaMissense 0.07, Benign/Likely benign, Cardiovascular phenotype; not specified; not provided
- A50S (p.Ala50Ser), rs28730751, ClinGen CA377553637, ClinVar RCV004519538, 1000Genomes rs28730751, AlphaMissense 0.07, MetaLR 0.11, Uncertain significance, Cardiovascular phenotype
- H51Y (p.His51Tyr), rs1554827989, ClinGen CA377553616, ClinVar RCV000624226, Ensembl rs1554827989, AlphaMissense 0.07, MetaLR 0.20, Uncertain significance, not specified
- P52A (p.Pro52Ala), rs397517248, ClinGen CA5598832, ClinVar RCV000250440, ClinVar RCV000694428, REVEL 0.29, CADD 6.72, Uncertain significance, Cardiovascular phenotype; Cardiomyopathy; ANKRD1-related dilated cardiomyopathy
- P52L (p.Pro52Leu), gnomAD rs1443210840, REVEL 0.11, CADD 4.27, Uncertain significance
- P52R (p.Pro52Arg), rs1443210840, ClinGen CA377553587, ClinVar RCV001962518, gnomAD rs1443210840, REVEL 0.07, CADD 3.01, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- P52S (p.Pro52Ser), rs397517248, ClinGen CA136823, ClinVar RCV000038844, ClinVar RCV002399382, REVEL 0.07, CADD 8.79, Conflicting interpretations, Cardiovascular phenotype; not specified; ANKRD1-related dilated cardiomyopathy
- P52T (p.Pro52Thr), ExAC rs397517248, TOPMed rs397517248, gnomAD rs397517248, REVEL 0.07, CADD 9.04, Likely benign
- T54S (p.Thr54Ser), Ensembl rs2120273676, REVEL 0.12, CADD 15.40
- L55P (p.Leu55Pro), rs1015674118, ClinGen CA211425683, ClinVar RCV003856875, TOPMed rs1015674118, REVEL 0.34, CADD 16.10, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- G56V (p.Gly56Val), rs2492962577, ClinGen CA377553505, ClinVar RCV002414530, Uncertain significance, Cardiovascular phenotype
- E57* (p.Glu57Ter), Ensembl rs2120273641
- E57G (p.Glu57Gly), gnomAD rs1342422889, REVEL 0.06, CADD 23.20
- Q58* (p.Gln58Ter), rs1290627165, ClinGen CA377553476, ClinVar RCV003829707, gnomAD rs1290627165, CADD 36.00, Uncertain significance
- Q58H (p.Gln58His), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- Q58K (p.Gln58Lys), gnomAD rs1290627165, REVEL 0.03, CADD 13.80, Uncertain significance
- Q59* (p.Gln59Ter), rs1057521825, ClinGen CA377553442, ClinVar RCV002401645, TOPMed rs1057521825, CADD 38.00, Uncertain significance
- Q59E (p.Gln59Glu), rs1057521825, ClinGen CA16606114, ClinVar RCV000422029, ClinVar RCV002402154, REVEL 0.10, CADD 16.70, Uncertain significance, not provided; ANKRD1-related dilated cardiomyopathy; Cardiovascular phenotype
- W60* (p.Trp60Ter), rs760365338, ClinGen CA335067, ClinVar RCV000802108, ClinVar RCV002408805, CADD 36.00, Uncertain significance
- W60R (p.Trp60Arg), rs2492962547, ClinGen CA377553420, ClinVar RCV003382135, Uncertain significance, Cardiovascular phenotype
- K61E (p.Lys61Glu), rs775086759, ClinGen CA5598827, ClinVar RCV000498944, ClinVar RCV003766806, REVEL 0.06, CADD 10.60, Uncertain significance, ANKRD1-related dilated cardiomyopathy; not provided
- K61N (p.Lys61Asn), rs2120273603, ClinGen CA377553372, ClinVar RCV001757104, Ensembl rs2120273603, REVEL 0.06, CADD 21.80, Uncertain significance, not provided
- S62R (p.Ser62Arg), ExAC rs766962252, TOPMed rs766962252, gnomAD rs766962252, REVEL 0.06, CADD 0.39, Likely benign
- S62T (p.Ser62Thr), Ensembl rs2120273598
- E63D (p.Glu63Asp), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
- E63K (p.Glu63Lys), rs143588078, ClinGen CA5598825, ClinVar RCV001372101, ClinVar RCV002413893, REVEL 0.22, CADD 22.70, Uncertain significance, Cardiovascular phenotype; not provided; ANKRD1-related dilated cardiomyopathy
- K64* (p.Lys64Ter), NCI-TCGA TCGA novel, Variant assessed as somatic; high impact.
- K64T (p.Lys64Thr), rs2120273578, ClinGen CA377553306, ClinVar RCV001905231, Ensembl rs2120273578, AlphaMissense 0.15, MetaLR 0.19, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- Q65* (p.Gln65Ter), ESP rs139169078, TOPMed rs139169078, gnomAD rs139169078, Likely benign
- Q65K (p.Gln65Lys), rs139169078, ClinGen CA211425666, ClinVar RCV001044105, ClinVar RCV001569814, REVEL 0.05, CADD 16.20, Conflicting interpretations, not specified; not provided; ANKRD1-related dilated cardiomyopathy
- Q65P (p.Gln65Pro), rs759803899, ClinGen CA5598824, ClinVar RCV000521563, ClinVar RCV002420320, REVEL 0.26, CADD 22.60, Uncertain significance, Cardiovascular phenotype; not provided; ANKRD1-related dilated cardiomyopathy
- R66* (p.Arg66Ter), rs397517249, ClinGen CA5598823, ClinVar RCV003529179, ClinVar RCV006343024, CADD 37.00, Benign
- R66G (p.Arg66Gly), rs397517249, ClinGen CA136826, ClinVar RCV000038845, ClinVar RCV000588271, REVEL 0.27, CADD 21.80, Benign/Likely benign, Cardiovascular phenotype; not specified; not provided
- R66Q (p.Arg66Gln), rs150797476, ClinGen CA136829, ClinVar RCV000038846, ClinVar RCV000172518, REVEL 0.29, CADD 22.10, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- E67D (p.Glu67Asp), Ensembl rs1589510717
- E67Q (p.Glu67Gln), TOPMed rs945448907, gnomAD rs945448907, REVEL 0.07, CADD 22.10
- A68G (p.Ala68Gly), rs2492962490, ClinGen CA377553248, ClinVar RCV004120701, Uncertain significance, Cardiovascular phenotype
- A68T (p.Ala68Thr), rs200249746, ClinGen CA237040, ClinVar RCV000171874, gnomAD rs200249746, REVEL 0.10, CADD 22.00, Uncertain significance, not provided
- E69D (p.Glu69Asp), TOPMed rs1847419797, gnomAD rs1847419797, REVEL 0.18, CADD 33.00
- E69K (p.Glu69Lys), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
- K72E (p.Lys72Glu), rs1564574800, ClinGen CA377553076, ClinVar RCV000701748, ClinVar RCV002424690, REVEL 0.18, CADD 22.90, Uncertain significance, Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- K72N (p.Lys72Asn), rs1847407710, ClinGen CA377553064, NCI-TCGA Cosmic COSV6331, ClinVar RCV001315490, AlphaMissense 0.36, MetaLR 0.18, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- K73E (p.Lys73Glu), rs1302708705, ClinGen CA377553059, ClinVar RCV002432865, gnomAD rs1302708705, REVEL 0.15, CADD 23.30, Uncertain significance, Cardiovascular phenotype
- K74N (p.Lys74Asn), rs1403366948, ClinGen CA377553031, ClinVar RCV002428199, TOPMed rs1403366948, REVEL 0.13, CADD 23.40, Uncertain significance, Cardiovascular phenotype
- E76I (p.Glu76Ile), rs1847407360, ClinGen CA916081613, ClinVar RCV001045721, Ensembl rs1847407360, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- E76K (p.Glu76Lys), gnomAD rs1400563129
- Q77E (p.Gln77Glu), rs869025362, ClinGen CA351967, ClinVar RCV000208357, Ensembl rs869025362, AlphaMissense 0.08, MetaLR 0.14, Uncertain significance
- Q77R (p.Gln77Arg), gnomAD rs1847407241, REVEL 0.07, CADD 22.10
- R78S (p.Arg78Ser), rs141376679, ClinGen CA175250, ClinVar RCV000150160, ClinVar RCV000560866, REVEL 0.43, CADD 25.40, Uncertain significance, Cardiovascular phenotype; not specified; ANKRD1-related dilated cardiomyopathy
- S79L (p.Ser79Leu), 1000Genomes rs2120272016, REVEL 0.24, CADD 22.70
- S79T (p.Ser79Thr), rs1028976027, ClinGen CA211424909, ClinVar RCV003529525, gnomAD rs1028976027, REVEL 0.07, CADD 21.90, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- K80N (p.Lys80Asn), rs1472596628, ClinGen CA377552948, ClinVar RCV003642511, gnomAD rs1472596628, REVEL 0.17, CADD 23.20, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- L81P (p.Leu81Pro), gnomAD rs1196778268, REVEL 0.53, CADD 29.70
- L81V (p.Leu81Val), gnomAD rs1428027802, REVEL 0.14, CADD 26.30, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- N83T (p.Asn83Thr), TOPMed rs1847406936
- E85D (p.Glu85Asp), TOPMed rs1453316775, gnomAD rs1453316775, REVEL 0.11, CADD 17.90
- D86E (p.Asp86Glu), TOPMed rs1445123382, gnomAD rs1445123382, REVEL 0.32, CADD 23.70, Likely benign
- D86G (p.Asp86Gly), ExAC rs759101459, gnomAD rs759101459, REVEL 0.42, CADD 28.00, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- D86H (p.Asp86His), rs573892607, ClinGen CA175247, ClinVar RCV000150159, ClinVar RCV001417860, REVEL 0.41, CADD 32.00, Conflicting interpretations, Cardiovascular phenotype; not specified; ANKRD1-related dilated cardiomyopathy
- L87F (p.Leu87Phe), ExAC rs751134864, gnomAD rs751134864, REVEL 0.40, CADD 28.60
- L87H (p.Leu87His), ExAC rs765783499, gnomAD rs765783499, REVEL 0.51, CADD 29.80, Uncertain significance, ANKRD1-related dilated cardiomyopathy; Cardiovascular phenotype
- I90L (p.Ile90Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- I90N (p.Ile90Asn), rs2492961103, ClinGen CA377552811, ClinVar RCV002437381, Uncertain significance, Cardiovascular phenotype
- I91T (p.Ile91Thr), rs1847406250, ClinGen CA377552794, ClinVar RCV002914192, Ensembl rs1847406250, REVEL 0.34, CADD 24.10, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- I91V (p.Ile91Val), rs773244166, ClinGen CA5598804, ClinVar RCV002437465, ExAC rs773244166, REVEL 0.07, CADD 16.60, Uncertain significance, Cardiovascular phenotype
- K94T (p.Lys94Thr), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- K95R (p.Lys95Arg), ExAC rs769732769
- R96K (p.Arg96Lys), gnomAD rs1294402907, REVEL 0.04, CADD 17.80
- R96M (p.Arg96Met), gnomAD rs1294402907, REVEL 0.21, CADD 25.00
- R100K (p.Arg100Lys), rs866997710, ClinGen CA211424881, ClinVar RCV002435585, ClinVar RCV005255719, REVEL 0.05, CADD 12.50, Conflicting interpretations, Cardiovascular phenotype; not provided
- R100S (p.Arg100Ser), rs1323094013, ClinGen CA377552494, ClinVar RCV000654869, ClinVar RCV002440393, REVEL 0.05, CADD 23.20, Uncertain significance, ANKRD1-related dilated cardiomyopathy; Cardiovascular phenotype
- P105L (p.Pro105Leu), rs1847405739, ClinGen CA377552460, ClinVar RCV001946243, TOPMed rs1847405739, REVEL 0.23, CADD 23.30, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- P105S (p.Pro105Ser), rs148189486, ClinGen CA249989, ClinVar RCV000172517, ClinVar RCV000622147, REVEL 0.37, CADD 20.60, Conflicting interpretations, Cardiovascular phenotype; not provided; ANKRD1-related dilated cardiomyopathy
- V106I (p.Val106Ile), rs201056963, ClinGen CA237037, ClinVar RCV000171873, ClinVar RCV004992048, REVEL 0.03, CADD 6.37, Conflicting interpretations, Cardiovascular phenotype; not provided
- V107A (p.Val107Ala), NCI-TCGA Cosmic COSV1007, REVEL 0.07, CADD 4.75, Variant assessed as somatic; moderate impact.
- V107L (p.Val107Leu), rs114435632, ClinGen CA136833, ClinVar RCV000038848, ClinVar RCV000172740, REVEL 0.13, CADD 7.64, Benign/Likely benign, Cardiovascular phenotype; not specified; not provided
- K108N (p.Lys108Asn), TOPMed rs1847405537, NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- E109D (p.Glu109Asp), Ensembl rs1847405508, Likely benign
- P110Q (p.Pro110Gln), gnomAD rs1477558904, REVEL 0.35, CADD 25.40, Uncertain significance, Cardiovascular phenotype
- P110S (p.Pro110Ser), rs200061926, ClinGen CA237034, ClinVar RCV000171872, ClinVar RCV001852084, REVEL 0.30, CADD 22.50, Uncertain significance, Cardiovascular phenotype; not provided; ANKRD1-related dilated cardiomyopathy
- P110T (p.Pro110Thr), rs200061926, ClinGen CA377552433, ClinVar RCV002742046, REVEL 0.30, CADD 22.20, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- P112H (p.Pro112His), NCI-TCGA TCGA novel, REVEL 0.29, CADD 24.70, Variant assessed as somatic; moderate impact.
- P112R (p.Pro112Arg), rs2492960991, ClinGen CA377552416, ClinVar RCV004107500, Uncertain significance, Cardiovascular phenotype
- E113* (p.Glu113Ter), rs183324142, ClinGen CA5598800, ClinVar RCV003296218, ClinVar RCV005422291, AlphaMissense 0.10, MetaLR 0.18, Uncertain significance
- E113K (p.Glu113Lys), rs183324142, ClinGen CA377552414, ClinVar RCV001315588, 1000Genomes rs183324142, AlphaMissense 0.10, MetaLR 0.18, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- I114N (p.Ile114Asn), Ensembl rs1564574731, REVEL 0.06, CADD 21.60
- I115T (p.Ile115Thr), rs886973409, ClinGen CA211424823, ClinVar RCV004519539, TOPMed rs886973409, REVEL 0.16, CADD 23.00, Uncertain significance, Cardiovascular phenotype
- T116A (p.Thr116Ala), rs774406553, ExAC rs774406553, gnomAD rs774406553, REVEL 0.04, CADD 17.30, Uncertain significance
- T116K (p.Thr116Lys), NCI-TCGA Cosmic COSV6331, REVEL 0.14, CADD 22.60, Uncertain significance
- T116M (p.Thr116Met), rs142354133, ClinGen CA5598747, NCI-TCGA Cosmic COSV6331, ClinVar RCV000215173, REVEL 0.26, CADD 24.90, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- E117K (p.Glu117Lys), rs1847400805, ClinGen CA377552379, ClinVar RCV004413437, gnomAD rs1847400805, REVEL 0.14, CADD 24.60, Uncertain significance, Cardiovascular phenotype
- P118T (p.Pro118Thr), gnomAD rs1382512098, REVEL 0.12, CADD 21.70, Uncertain significance, Cardiovascular phenotype
- D120H (p.Asp120His), rs778238821, ClinGen CA377552359, ClinVar RCV003529206, ClinVar RCV006343027, REVEL 0.45, CADD 28.40, Uncertain significance, ANKRD1-related dilated cardiomyopathy; Cardiovascular phenotype
- D120N (p.Asp120Asn), ExAC rs778238821, TOPMed rs778238821, gnomAD rs778238821, Uncertain significance
- V121A (p.Val121Ala), Ensembl rs997524452
- P122A (p.Pro122Ala), rs756392442, ClinGen CA5598745, ClinVar RCV000705569, ClinVar RCV002458313, REVEL 0.04, AlphaMissense 0.08, Conflicting interpretations, not provided; ANKRD1-related dilated cardiomyopathy; Cardiovascular phenotype
- P122L (p.Pro122Leu), ExAC rs746696408, gnomAD rs746696408, REVEL 0.15, CADD 23.00
- P122S (p.Pro122Ser), rs756392442, ClinGen CA377552346, ClinVar RCV002731631, ExAC rs756392442, AlphaMissense 0.08, MetaLR 0.12, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- T123K (p.Thr123Lys), rs145387010, ClinGen CA377552340, ClinVar RCV002049380, 1000Genomes rs145387010, AlphaMissense 0.09, MetaLR 0.14, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- T123M (p.Thr123Met), rs145387010, ClinGen CA245339, ClinVar RCV000171828, ClinVar RCV000183297, REVEL 0.35, AlphaMissense 0.09, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- F124L (p.Phe124Leu), ExAC rs750012924, TOPMed rs750012924, gnomAD rs750012924, REVEL 0.44, CADD 26.50
- A127P (p.Ala127Pro), gnomAD rs1166773924, REVEL 0.76, CADD 27.30
- A128S (p.Ala128Ser), rs887010560, ClinGen CA211424319, ClinVar RCV004138921, Ensembl rs887010560, REVEL 0.41, CADD 25.40, Uncertain significance, Cardiovascular phenotype
- L129V (p.Leu129Val), TOPMed rs1243121367, gnomAD rs1243121367, REVEL 0.04, CADD 16.50, Uncertain significance, Cardiovascular phenotype
- E130* (p.Glu130Ter), rs1048316962, ClinGen CA211424309, ClinVar RCV000618783, ClinVar RCV000770305, CADD 40.00, Uncertain significance
- E130V (p.Glu130Val), rs1321608531, ClinGen CA377552296, ClinVar RCV002640559, TOPMed rs1321608531, AlphaMissense 0.46, MetaLR 0.32, Uncertain significance, ANKRD1-related dilated cardiomyopathy
- P134S (p.Pro134Ser), rs370001020, ClinGen CA5598742, ClinVar RCV002375708, ClinVar RCV006470655, REVEL 0.05, CADD 22.40, Uncertain significance, Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- V135A (p.Val135Ala), rs995351186, ClinGen CA377552230, NCI-TCGA Cosmic COSV6331, ClinVar RCV004519540, AlphaMissense 0.44, MetaLR 0.37, Uncertain significance, Cardiovascular phenotype
- V135E (p.Val135Glu), rs995351186, ClinGen CA211424298, ClinVar RCV000815319, ClinVar RCV002325601, REVEL 0.68, AlphaMissense 0.44, Uncertain significance, Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- V136A (p.Val136Ala), rs1208266830, ClinGen CA377552220, ClinVar RCV001346089, ClinVar RCV004995698, REVEL 0.35, CADD 24.80, Uncertain significance, Cardiovascular phenotype; ANKRD1-related dilated cardiomyopathy
- K138E (p.Lys138Glu), Ensembl rs1564574554
- F139L (p.Phe139Leu), rs201398260, ClinGen CA136841, ClinVar RCV000038852, ClinVar RCV000767133, REVEL 0.20, CADD 26.30, Conflicting interpretations, Cardiovascular phenotype; not specified; not provided
- F139V (p.Phe139Val), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
- F139Y (p.Phe139Tyr), NCI-TCGA Cosmic COSV6331, Variant assessed as somatic; moderate impact.
Public ANKRD1 analysis runs
- ANKRD1 analysis run — ANKRD1 (605 variants) — completed 2026-08-21