ABCG5 (Q9H222) variants and mutations
ABCG5 (also known as Q9H222) is a human protein-coding gene encoding an ATP-binding cassette sub-family G member 5 protein. Together with ABCG8, it limits sterol accumulation by promoting cholesterol and plant-sterol excretion into bile and back into the intestinal lumen. Biallelic loss-of-function variants cause sitosterolemia, with elevated plant sterols, premature atherosclerosis, and sometimes hematologic abnormalities. This analysis covers 1,285 ABCG5 variants and mutations. Of these, 86% have computational variant effect predictions. Disease context includes sitosterolemia, sitosterolemia 2, and cholelithiasis. Example ABCG5 variants include M1T, M1V, and G2C.
Variant analysis overview
- Gene: ABCG5
- Protein: Q9H222
- UniProt accession: Q9H222
- Organism: Homo sapiens
- Variants analyzed: 1285
- Variant scope: all variants
- Completed: 2026-08-20
Variant and mutation evidence
- Variant composition: 1,026 unspecified-consequence records; 18 frameshift variants; 108 synonymous variants; 120 missense variants; 3 stop-gained variants; 5 splice-region variants; 1 in-frame insertions; 4 substitution
- Prediction scores: 1,107 variants have prediction scores (86% of the analyzed set).
Clinical, disease, and population context
- Disease context: 25 disease associations are represented. Top associations: sitosterolemia, sitosterolemia 2, cholelithiasis, sitosterolemia 1, Abnormality of the cardiovascular system, Disorder of lipid metabolism, metabolic disease, Hypercholesterolemia, gallstones, Cholecystitis, familial hypercholesterolemia, gallbladder disorder.
Protein structure and variant hotspots
- Protein features: 6 transmembrane segments; 2 domains; 1 binding sites; 2 post-translational modification sites.
- Structural context: 1,021 variants have structural context.
- PTM context: 4 variants overlap post-translational modification sites.
Data sources
Evidence in this analysis draws on EBI Proteins Variation, UniProt, gnomAD v4, EuropePMC, 3D Hotspot Analysis, Interaction Network Analysis, Protein Data Bank, AlphaFold DB, gnomAD constraint, Open Targets, ClinGen, MaveDB, LitVar.
Notable ABCG5 variants
Examples include M1T, M1V, G2C, G2V, D3E, D3N, D3V, L4F. Listed records include available protein-change notation, database identifiers, clinical classifications, computational predictions, population evidence, experimental measurements, and disease context.
- M1T (p.Met1Thr), rs745785626, ClinGen CA1636826, ClinVar RCV001346003, MetaLR 0.59, MetaSVM 0.22, Conflicting interpretations, Sitosterolemia 1; not provided
- M1V (p.Met1Val), rs755998551, ClinGen CA1636827, ClinVar RCV003612382, MetaLR 0.56, MetaSVM -0.02, Uncertain significance, Sitosterolemia
- G2C (p.Gly2Cys), cosmic curated COSV99575
- G2V (p.Gly2Val), Ensembl rs1668440469, SIFT 0.04
- D3E (p.Asp3Glu), Ensembl rs1572811782
- D3N (p.Asp3Asn), NCI-TCGA Cosmic COSV9957, cosmic curated COSV99575, Ensembl rs1668440341, SIFT 1.00, Variant assessed as somatic; moderate impact.
- D3V (p.Asp3Val), 1000Genomes rs575118638, CADD 16.00
- L4F (p.Leu4Phe), ExAC rs751275236, TOPMed rs751275236, gnomAD rs751275236, CADD 7.20, PolyPhen-2 0.00, Uncertain significance, Cardiovascular phenotype
- L4I (p.Leu4Ile), rs751275236, ClinGen CA1636823, NCI-TCGA Cosmic COSV5321, cosmic curated COSV53211, CADD 11.50, PolyPhen-2 0.00, Uncertain significance, Cardiovascular phenotype
- S5L (p.Ser5Leu), Ensembl rs1668439625, SIFT 0.51, Uncertain significance, Sitosterolemia 2
- S6C (p.Ser6Cys), cosmic curated COSV53212, gnomAD rs1315307010, CADD 0.42, PolyPhen-2 0.00
- S6F (p.Ser6Phe), cosmic curated COSV10502, CADD 0.14, PolyPhen-2 0.00
- L7F (p.Leu7Phe), cosmic curated COSV10807, CADD 4.97, PolyPhen-2 0.09
- L7S (p.Leu7Ser), cosmic curated COSV10502
- L7V (p.Leu7Val), cosmic curated COSV10502
- T8A (p.Thr8Ala), gnomAD rs1668439161, CADD 4.82, PolyPhen-2 0.00
- T8I (p.Thr8Ile), ExAC rs757846931, TOPMed rs757846931, gnomAD rs757846931, CADD 3.05, PolyPhen-2 0.00, Uncertain significance, Sitosterolemia 2
- T8N (p.Thr8Asn), rs757846931, ClinGen CA346662163, ClinVar RCV001136900, ExAC rs757846931, CADD 6.80, PolyPhen-2 0.02, Uncertain significance, Sitosterolemia 1
- T8S (p.Thr8Ser), ExAC rs757846931, TOPMed rs757846931, gnomAD rs757846931, SIFT 0.54, Uncertain significance
- P9L (p.Pro9Leu), NCI-TCGA Cosmic COSV5321, cosmic curated COSV53213, SIFT 0.21, Variant assessed as somatic; moderate impact.
- P9T (p.Pro9Thr), rs1301882747, ClinGen CA346662153, ClinVar RCV002426223, TOPMed rs1301882747, CADD 4.92, PolyPhen-2 0.00, Uncertain significance, Cardiovascular phenotype
- G10* (p.Gly10Ter), NCI-TCGA Cosmic COSV5321, Variant assessed as somatic; high impact.
- G10R (p.Gly10Arg), rs761311404, ExAC rs761311404, TOPMed rs761311404, gnomAD rs761311404, CADD 0.00, PolyPhen-2 0.00, Uncertain significance, Cardiovascular phenotype
- S12Y (p.Ser12Tyr), cosmic curated COSV99575
- M13I (p.Met13Ile), rs572875739, NCI-TCGA Cosmic COSV5321, NCI-TCGA Cosmic COSV9957, cosmic curated COSV99575, CADD 0.04, PolyPhen-2 0.00, Uncertain significance, not specified; Cardiovascular phenotype
- M13V (p.Met13Val), ExAC rs762253861
- G14C (p.Gly14Cys), NCI-TCGA Cosmic COSV9957, cosmic curated COSV99575, CADD 18.90, PolyPhen-2 0.54, Variant assessed as somatic; moderate impact.
- G14D (p.Gly14Asp), gnomAD rs1166674418, CADD 1.53, PolyPhen-2 0.00, Uncertain significance
- G14S (p.Gly14Ser), gnomAD rs1668437409, CADD 7.30, PolyPhen-2 0.06, Uncertain significance, not specified
- G14V (p.Gly14Val), gnomAD rs1166674418, CADD 2.93, PolyPhen-2 0.13, Uncertain significance, ABCG5-related disorder
- L15F (p.Leu15Phe), rs372312214, ClinGen CA346662072, ClinVar RCV002572686, cosmic curated COSV53213, AlphaMissense 0.07, MetaLR 0.46, Uncertain significance, Sitosterolemia
- L15I (p.Leu15Ile), rs372312214, ClinGen CA46426251, ClinVar RCV002571925, ESP rs372312214, AlphaMissense 0.07, MetaLR 0.46, Uncertain significance, Sitosterolemia
- L15V (p.Leu15Val), rs372312214, ClinGen CA1636812, ClinVar RCV000350361, ClinVar RCV002328782, AlphaMissense 0.07, MetaLR 0.46, Uncertain significance, Cardiovascular phenotype; Sitosterolemia; not provided
- Q16* (p.Gln16Ter), rs387906912, ClinGen CA259823, ClinVar RCV000023441, Ensembl rs387906912, Pathogenic
- V17E (p.Val17Glu), 1000Genomes rs72542427, ESP rs72542427, ExAC rs72542427, TOPMed rs72542427, CADD 0.02, PolyPhen-2 0.00, Likely benign
- V17G (p.Val17Gly), rs72542427, ClinGen CA1636811, ClinVar RCV000393828, ClinVar RCV000892629, CADD 0.04, PolyPhen-2 0.00, Conflicting interpretations, Sitosterolemia 2; not specified; Sitosterolemia
- V17L (p.Val17Leu), gnomAD rs1177967200, CADD 2.33, PolyPhen-2 0.00
- N18S (p.Asn18Ser), ExAC rs769836264, gnomAD rs769836264, CADD 2.91, PolyPhen-2 0.00
- R19I (p.Arg19Ile), 1000Genomes rs745875586, ExAC rs745875586, TOPMed rs745875586, gnomAD rs745875586, AlphaMissense 0.08, MetaLR 0.45, Uncertain significance, Cardiovascular phenotype
- R19K (p.Arg19Lys), rs745875586, ClinGen CA346662014, cosmic curated COSV53210, ClinVar RCV004418200, AlphaMissense 0.08, MetaLR 0.45, Uncertain significance, Cardiovascular phenotype
- G20D (p.Gly20Asp), Ensembl rs1668435842
- Q22* (p.Gln22Ter), rs781098379, ClinGen CA1636808, ClinVar RCV002282969, ClinVar RCV002283584, CADD 35.00, Pathogenic
- S23T (p.Ser23Thr), TOPMed rs1668435574, CADD 8.52, PolyPhen-2 0.00
- S24F (p.Ser24Phe), cosmic curated COSV53211, SIFT 0.01
- L25P (p.Leu25Pro), NCI-TCGA TCGA novel, TOPMed rs1668434997, gnomAD rs1668434997, CADD 12.10, PolyPhen-2 0.00, Variant assessed as somatic; moderate impact.
- L25V (p.Leu25Val), rs1668435149, ClinGen CA346661933, ClinVar RCV004171371, gnomAD rs1668435149, CADD 5.28, PolyPhen-2 0.02, Uncertain significance, Cardiovascular phenotype
- E26A (p.Glu26Ala), TOPMed rs1393088059
- E26D (p.Glu26Asp), rs144622073, ClinGen CA1636807, ClinVar RCV001136898, ClinVar RCV002418591, CADD 17.30, PolyPhen-2 0.04, Uncertain significance, Sitosterolemia 2; Sitosterolemia; Sitosterolemia 1
- E26G (p.Glu26Gly), TOPMed rs1393088059, CADD 17.50, PolyPhen-2 0.00
- E26K (p.Glu26Lys), cosmic curated COSV53211, Uncertain significance, Sitosterolemia 2
- G27A (p.Gly27Ala), rs56204478, ClinGen CA1636806, ClinVar RCV000384239, ClinVar RCV000852225, CADD 3.43, PolyPhen-2 0.00, Conflicting interpretations, Sitosterolemia 1; Cardiovascular phenotype; not specified
- G27E (p.Gly27Glu), 1000Genomes rs56204478, ESP rs56204478, ExAC rs56204478, TOPMed rs56204478, CADD 1.50, PolyPhen-2 0.00, Benign
- G27R (p.Gly27Arg), NCI-TCGA Cosmic COSV5321, cosmic curated COSV53210, CADD 11.30, Variant assessed as somatic; moderate impact.
- A28P (p.Ala28Pro), TOPMed rs980495592, gnomAD rs980495592, CADD 13.30, PolyPhen-2 0.09, Uncertain significance
- A28S (p.Ala28Ser), rs980495592, ClinGen CA346661892, ClinVar RCV002011244, TOPMed rs980495592, CADD 7.63, PolyPhen-2 0.02, Uncertain significance, Sitosterolemia
- P29L (p.Pro29Leu), rs1558783068, ClinGen CA346661875, ClinVar RCV000731163, gnomAD rs1558783068, CADD 5.71, Uncertain significance, not provided
- A30D (p.Ala30Asp), cosmic curated COSV99575, CADD 5.50, PolyPhen-2 0.04
- T31N (p.Thr31Asn), Ensembl rs1449635921
- T31P (p.Thr31Pro), Ensembl rs187767254
- A32T (p.Ala32Thr), rs758017120, ClinGen CA1636804, ClinVar RCV000503124, ExAC rs758017120, CADD 2.16, PolyPhen-2 0.00, Uncertain significance, not specified
- P33L (p.Pro33Leu), rs778605187, ClinGen CA1636803, ClinVar RCV002928691, ClinVar RCV005382502, CADD 4.40, PolyPhen-2 0.00, Conflicting interpretations, Cardiovascular phenotype; Sitosterolemia
- P33R (p.Pro33Arg), rs778605187, ClinGen CA1636802, ClinVar RCV000281113, ClinVar RCV002379142, CADD 2.73, PolyPhen-2 0.01, Uncertain significance, Sitosterolemia 2; Cardiovascular phenotype; not provided
- P33S (p.Pro33Ser), gnomAD rs1305650144
- E34D (p.Glu34Asp), gnomAD rs1295215814, CADD 8.40, PolyPhen-2 0.04
- E34K (p.Glu34Lys), cosmic curated COSV10502, Ensembl rs980942112
- P35L (p.Pro35Leu), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- P35S (p.Pro35Ser), gnomAD rs1456234754, SIFT 0.86
- H36P (p.His36Pro), Ensembl rs201992386
- H36Y (p.His36Tyr), Ensembl rs892316704, CADD 22.90, PolyPhen-2 0.59
- S37I (p.Ser37Ile), NCI-TCGA Cosmic COSV5321, cosmic curated COSV53213, SIFT 0.01, Variant assessed as somatic; moderate impact.
- L38V (p.Leu38Val), rs375829761, ClinGen CA1636800, ClinVar RCV000593479, ClinVar RCV001867979, CADD 17.20, PolyPhen-2 0.35, Uncertain significance, not specified; Cardiovascular phenotype; not provided
- G39D (p.Gly39Asp), rs371929020, ClinGen CA1636799, ClinVar RCV001307964, ClinVar RCV002327681, CADD 15.30, PolyPhen-2 0.16, Uncertain significance, Cardiovascular phenotype; not provided; Sitosterolemia 2
- G39S (p.Gly39Ser), gnomAD rs1159565661, CADD 2.94, PolyPhen-2 0.00
- L41V (p.Leu41Val), rs1030894919, ClinGen CA46426095, ClinVar RCV001761283, ClinVar RCV002540441, CADD 8.79, PolyPhen-2 0.03, Uncertain significance, not provided; Sitosterolemia; Cardiovascular phenotype
- A43D (p.Ala43Asp), rs1181566629, gnomAD rs1181566629, CADD 17.00, PolyPhen-2 0.05, Variant assessed as somatic; moderate impact.
- A43V (p.Ala43Val), gnomAD rs1181566629, CADD 7.36, PolyPhen-2 0.00, Likely benign, Cardiovascular phenotype
- S44A (p.Ser44Ala), TOPMed rs1001173239, gnomAD rs1001173239, CADD 24.10, PolyPhen-2 0.22, Likely pathogenic, Sitosterolemia
- S44F (p.Ser44Phe), cosmic curated COSV53212, 1000Genomes rs557687545, ExAC rs557687545, gnomAD rs557687545, CADD 27.00, PolyPhen-2 0.59
- Y45* (p.Tyr45Ter), ExAC rs763278758, TOPMed rs763278758, gnomAD rs763278758, CADD 37.00
- Y45H (p.Tyr45His), gnomAD rs1208543291, CADD 28.30, PolyPhen-2 0.84
- S46R (p.Ser46Arg), cosmic curated COSV53211, ExAC rs775574718, TOPMed rs775574718, gnomAD rs775574718, CADD 11.70, PolyPhen-2 0.67, Likely benign
- V47F (p.Val47Phe), rs72542426, ClinGen CA1636791, ClinVar RCV001136896, ClinVar RCV001512079, CADD 17.90, PolyPhen-2 0.48, Conflicting interpretations, Sitosterolemia 1; not provided; Sitosterolemia 2
- V47I (p.Val47Ile), rs72542426, ClinGen CA1636793, cosmic curated COSV53209, ClinVar RCV000731084, CADD 6.57, PolyPhen-2 0.00, Conflicting interpretations, Sitosterolemia 2; Sitosterolemia; Cardiovascular phenotype
- V47L (p.Val47Leu), rs72542426, ClinGen CA1636792, ClinVar RCV001136897, ClinVar RCV002393364, CADD 13.20, PolyPhen-2 0.05, Uncertain significance, Cardiovascular phenotype; Sitosterolemia 2; Sitosterolemia 1
- S48C (p.Ser48Cys), NCI-TCGA TCGA novel, Variant assessed as somatic; moderate impact.
- S48R (p.Ser48Arg), gnomAD rs1182768861, CADD 15.40
- S48T (p.Ser48Thr), TOPMed rs1668429557, CADD 25.90, PolyPhen-2 0.41
- R50C (p.Arg50Cys), rs6756629, ClinGen CA1636763, cosmic curated COSV53211, ClinVar RCV000272378, CADD 23.60, PolyPhen-2 0.65, Benign/Likely benign, not provided; Sitosterolemia; Cardiovascular phenotype
- R50G (p.Arg50Gly), 1000Genomes rs6756629, ESP rs6756629, ExAC rs6756629, TOPMed rs6756629, Benign
- R50H (p.Arg50His), rs200036521, ClinGen CA1636761, ClinVar RCV004418097, 1000Genomes rs200036521, CADD 3.37, PolyPhen-2 0.01, Uncertain significance, Cardiovascular phenotype
- R50L (p.Arg50Leu), rs200036521, ClinGen CA1636762, ClinVar RCV004517507, 1000Genomes rs200036521, CADD 9.93, PolyPhen-2 0.20, Uncertain significance, Cardiovascular phenotype
- R50P (p.Arg50Pro), 1000Genomes rs200036521, ExAC rs200036521, TOPMed rs200036521, gnomAD rs200036521, CADD 16.80, PolyPhen-2 0.52, Uncertain significance
- R50S (p.Arg50Ser), 1000Genomes rs6756629, ESP rs6756629, ExAC rs6756629, TOPMed rs6756629, Benign
- V51M (p.Val51Met), rs551349294, ClinGen CA1636759, cosmic curated COSV53210, ClinVar RCV001143475, CADD 20.30, PolyPhen-2 0.83, Uncertain significance, Cardiovascular phenotype; Sitosterolemia 1
- R52K (p.Arg52Lys), rs758798787, ClinGen CA346661622, cosmic curated COSV10502, ClinVar RCV004418116, CADD 20.00, PolyPhen-2 0.01, Uncertain significance, Cardiovascular phenotype
- R52M (p.Arg52Met), ExAC rs758798787, TOPMed rs758798787, gnomAD rs758798787, CADD 21.10, PolyPhen-2 0.11, Uncertain significance, Cardiovascular phenotype
- P53L (p.Pro53Leu), rs1395568891, ClinGen CA346661614, ClinVar RCV003306343, ClinVar RCV003420650, CADD 25.00, PolyPhen-2 0.73, Uncertain significance, ABCG5-related disorder; Cardiovascular phenotype; Sitosterolemia
- P53S (p.Pro53Ser), ESP rs372772883, ExAC rs372772883, TOPMed rs372772883, gnomAD rs372772883, CADD 22.20, PolyPhen-2 0.65
- P53T (p.Pro53Thr), ESP rs372772883, ExAC rs372772883, TOPMed rs372772883, gnomAD rs372772883
- W54* (p.Trp54Ter), gnomAD rs1371222213, CADD 40.00
- W55* (p.Trp55Ter), cosmic curated COSV10455
- W55R (p.Trp55Arg), Ensembl rs1668385451, SIFT 0.01
- D56A (p.Asp56Ala), ExAC rs765464603, SIFT 0.05, Uncertain significance, Cardiovascular phenotype
- I57V (p.Ile57Val), ESP rs144206840, TOPMed rs144206840, gnomAD rs144206840, CADD 0.00, PolyPhen-2 0.00, Uncertain significance, Cardiovascular phenotype
- T58P (p.Thr58Pro), NCI-TCGA Cosmic COSV5321, cosmic curated COSV53213, Variant assessed as somatic; moderate impact.
- S59F (p.Ser59Phe), gnomAD rs1428419912, CADD 23.00, PolyPhen-2 0.83, Uncertain significance, Cardiovascular phenotype
- R61G (p.Arg61Gly), ExAC rs766545187, TOPMed rs766545187, gnomAD rs766545187, CADD 6.45, PolyPhen-2 0.02, Uncertain significance
- R61L (p.Arg61Leu), ESP rs149599171, ExAC rs149599171, TOPMed rs149599171, gnomAD rs149599171, CADD 6.88, Uncertain significance
- R61P (p.Arg61Pro), ESP rs149599171, ExAC rs149599171, TOPMed rs149599171, gnomAD rs149599171, CADD 14.50, PolyPhen-2 0.11, Uncertain significance
- R61Q (p.Arg61Gln), rs149599171, ClinGen CA1636752, ClinVar RCV000362294, ClinVar RCV000523427, CADD 5.22, PolyPhen-2 0.00, Uncertain significance, not provided; Sitosterolemia 2; Sitosterolemia 1
- R61W (p.Arg61Trp), rs766545187, ClinGen CA1636753, ClinVar RCV000734914, ClinVar RCV001343394, CADD 7.65, PolyPhen-2 0.00, Uncertain significance, Sitosterolemia; Cardiovascular phenotype; not provided
- Q62R (p.Gln62Arg), rs1184914797, ClinGen CA346661555, ClinVar RCV003324225, ClinVar RCV004985331, CADD 12.00, PolyPhen-2 0.00, Uncertain significance, not specified; Cardiovascular phenotype
- Q63* (p.Gln63Ter), TOPMed rs986977157, gnomAD rs986977157, CADD 35.00
- Q63P (p.Gln63Pro), cosmic curated COSV53212
- W64* (p.Trp64Ter), cosmic curated COSV53213, cosmic curated COSV53210, CADD 38.00
- W64G (p.Trp64Gly), TOPMed rs1302886563
- T65N (p.Thr65Asn), ExAC rs773214529, TOPMed rs773214529, gnomAD rs773214529, CADD 10.40, PolyPhen-2 0.00
- R66K (p.Arg66Lys), gnomAD rs1668383501, CADD 18.60, PolyPhen-2 0.02, Uncertain significance, Cardiovascular phenotype
- Q67E (p.Gln67Glu), NCI-TCGA Cosmic COSV5321, cosmic curated COSV53211, Variant assessed as somatic; moderate impact.
- I68F (p.Ile68Phe), TOPMed rs1403673533, gnomAD rs1403673533, CADD 24.00, PolyPhen-2 0.73, Uncertain significance, Cardiovascular phenotype
- L69R (p.Leu69Arg), gnomAD rs1668383231, CADD 26.90
- K70E (p.Lys70Glu), TOPMed rs1668382922, CADD 23.30, PolyPhen-2 0.39
- K70T (p.Lys70Thr), gnomAD rs1668382783, CADD 23.60
- D71E (p.Asp71Glu), ExAC rs774338179, TOPMed rs774338179, gnomAD rs774338179, CADD 2.27, PolyPhen-2 0.17, Uncertain significance, Cardiovascular phenotype; not provided
- D71G (p.Asp71Gly), rs761690671, ClinGen CA1636749, ClinVar RCV002417742, ExAC rs761690671, CADD 25.50, PolyPhen-2 0.94, Uncertain significance, Cardiovascular phenotype
- D71H (p.Asp71His), ExAC rs767291426, gnomAD rs767291426, CADD 23.60, PolyPhen-2 0.98
- D71N (p.Asp71Asn), ExAC rs767291426, gnomAD rs767291426, CADD 23.50, PolyPhen-2 0.91
- V72A (p.Val72Ala), ExAC rs749017748, TOPMed rs749017748, gnomAD rs749017748, CADD 23.00, PolyPhen-2 0.28
- V72I (p.Val72Ile), rs768541576, ClinGen CA1636747, NCI-TCGA Cosmic COSV5320, cosmic curated COSV53209, CADD 14.00, PolyPhen-2 0.01, Uncertain significance, Cardiovascular phenotype
- S73F (p.Ser73Phe), cosmic curated COSV53210
- S73Y (p.Ser73Tyr), Ensembl rs948272335
- L74F (p.Leu74Phe), NCI-TCGA TCGA novel, CADD 8.36, PolyPhen-2 0.01, Variant assessed as somatic; moderate impact.
- L74V (p.Leu74Val), rs775270938, ClinGen CA1636745, ClinVar RCV000733169, ExAC rs775270938, CADD 15.60, PolyPhen-2 0.27, Uncertain significance, not provided
- Y75* (p.Tyr75Ter), ExAC rs745310708, TOPMed rs745310708, gnomAD rs745310708, CADD 33.00, Likely benign
- Y75C (p.Tyr75Cys), ExAC rs769363958, TOPMed rs769363958, gnomAD rs769363958, CADD 23.70, PolyPhen-2 0.63
- Y75D (p.Tyr75Asp), gnomAD rs1282693864, CADD 23.20, PolyPhen-2 0.29, Uncertain significance, Cardiovascular phenotype
- Y75H (p.Tyr75His), gnomAD rs1282693864, CADD 17.40, PolyPhen-2 0.00, Uncertain significance, Cardiovascular phenotype
- Y75S (p.Tyr75Ser), ExAC rs769363958, TOPMed rs769363958, gnomAD rs769363958, CADD 18.40, PolyPhen-2 0.15
- V76A (p.Val76Ala), NCI-TCGA Cosmic COSV9957, cosmic curated COSV99575, Variant assessed as somatic; moderate impact.
- V76L (p.Val76Leu), rs368811625, ClinGen CA346661468, ClinVar RCV002443875, AlphaMissense 0.10, MetaLR 0.69, Uncertain significance, Cardiovascular phenotype
- V76M (p.Val76Met), rs368811625, ClinGen CA1636742, ClinVar RCV001062708, ClinVar RCV002445326, AlphaMissense 0.10, MetaLR 0.69, Uncertain significance, Cardiovascular phenotype; Sitosterolemia
- E77* (p.Glu77Ter), rs119480070, ClinGen CA253377, ClinVar RCV000005269, ExAC rs119480070, CADD 38.00, Pathogenic
- S78I (p.Ser78Ile), TOPMed rs1257853786, gnomAD rs1257853786, CADD 24.90, PolyPhen-2 0.95
- S78N (p.Ser78Asn), TOPMed rs1257853786, gnomAD rs1257853786, CADD 24.30, PolyPhen-2 0.86
- S78R (p.Ser78Arg), rs748628439, NCI-TCGA Cosmic COSV5320, cosmic curated COSV53209, CADD 13.00, PolyPhen-2 0.97, Likely benign
- S78T (p.Ser78Thr), TOPMed rs1257853786, gnomAD rs1257853786, CADD 24.10
- G79R (p.Gly79Arg), rs142125966, ClinGen CA1636740, ClinVar RCV000734930, ClinVar RCV001143473, CADD 25.00, PolyPhen-2 1.00, Uncertain significance, Sitosterolemia; Sitosterolemia 1; Cardiovascular phenotype
- G79V (p.Gly79Val), gnomAD rs1668379427, CADD 23.70
- Q80* (p.Gln80Ter), cosmic curated COSV99575
- Q80K (p.Gln80Lys), rs373819340, ClinGen CA1636739, ClinVar RCV001873908, ClinVar RCV002261396, CADD 22.90, PolyPhen-2 0.27, Uncertain significance, Sitosterolemia 2; Sitosterolemia; not provided
- I81M (p.Ile81Met), ExAC rs766455908, TOPMed rs766455908, gnomAD rs766455908, CADD 15.30, PolyPhen-2 0.36, Uncertain significance, Cardiovascular phenotype
- I81T (p.Ile81Thr), rs1441999437, ClinGen CA346661433, ClinVar RCV002459877, ClinVar RCV003101808, CADD 20.70, PolyPhen-2 0.01, Uncertain significance, Cardiovascular phenotype; Sitosterolemia
- M82T (p.Met82Thr), ExAC rs756224121, gnomAD rs756224121, REVEL 0.66, CADD 21.90
- C83* (p.Cys83Ter), NCI-TCGA TCGA novel, CADD 37.00, Variant assessed as somatic; high impact.
- I84L (p.Ile84Leu), cosmic curated COSV53212
- I84V (p.Ile84Val), TOPMed rs1418182935, gnomAD rs1418182935, REVEL 0.16, CADD 25.10, Uncertain significance, Sitosterolemia
- L85R (p.Leu85Arg), TOPMed rs1668377745, REVEL 0.75, CADD 24.60
- L85V (p.Leu85Val), TOPMed rs1668377892, REVEL 0.68, CADD 5.82
- G86E (p.Gly86Glu), cosmic curated COSV53209
- S87I (p.Ser87Ile), rs1471323186, ClinGen CA346661391, ClinVar RCV003306344, TOPMed rs1471323186, REVEL 0.69, CADD 24.60, Uncertain significance, Cardiovascular phenotype
- S87N (p.Ser87Asn), TOPMed rs1471323186, gnomAD rs1471323186, REVEL 0.38, CADD 16.70, Uncertain significance
- S87R (p.Ser87Arg), TOPMed rs1232276390, gnomAD rs1232276390, REVEL 0.67, CADD 24.70
- S88* (p.Ser88Ter), ExAC rs767611945, TOPMed rs767611945, gnomAD rs767611945, CADD 43.00
- G89A (p.Gly89Ala), rs886056031, ClinGen CA10613855, ClinVar RCV000307666, gnomAD rs886056031, REVEL 0.85, CADD 27.20, Uncertain significance, Sitosterolemia 1
- G89D (p.Gly89Asp), gnomAD rs886056031, REVEL 0.94, CADD 32.00, Uncertain significance
- G89S (p.Gly89Ser), TOPMed rs1453206674, gnomAD rs1453206674, REVEL 0.81, CADD 34.00
- S90A (p.Ser90Ala), TOPMed rs1476302309
- S90C (p.Ser90Cys), gnomAD rs1176174466
- S90F (p.Ser90Phe), gnomAD rs1176174466, MetaLR 0.93, MetaSVM 1.08
- G91E (p.Gly91Glu), rs749587717, ClinGen CA1636718, ClinVar RCV002245434, ExAC rs749587717, REVEL 0.97, CADD 26.90, Uncertain significance, Sitosterolemia 1
- G91R (p.Gly91Arg), TOPMed rs902259474, gnomAD rs902259474, REVEL 0.93, CADD 24.60, Uncertain significance, Cardiovascular phenotype
- K92E (p.Lys92Glu), rs2466095732, ClinGen CA346668321, ClinVar RCV003055204, REVEL 0.86, CADD 29.80, Uncertain significance, Sitosterolemia
- K92N (p.Lys92Asn), gnomAD rs1172899550, REVEL 0.62, CADD 22.30
- T94M (p.Thr94Met), rs558993616, ClinGen CA346668290, ClinVar RCV001143472, ExAC rs558993616, REVEL 0.77, CADD 32.00, Uncertain significance, Sitosterolemia 1
- T94R (p.Thr94Arg), rs558993616, ClinGen CA1636717, ClinVar RCV000275956, ClinVar RCV001094755, REVEL 0.76, CADD 31.00, Uncertain significance, Sitosterolemia 1; Cardiovascular phenotype; not provided
- L96R (p.Leu96Arg), gnomAD rs1667984526
- A98C (p.Ala98Cys), rs1667984117, ClinGen CA2493937548, ClinVar RCV001329275, ClinVar RCV003135984, Uncertain significance, Sitosterolemia 1; Sitosterolemia 2; Sitosterolemia
- A98G (p.Ala98Gly), rs145164937, ClinGen CA1636713, ClinVar RCV000376941, ClinVar RCV000766455, REVEL 0.87, CADD 29.80, Conflicting interpretations, Cardiovascular phenotype; Sitosterolemia 1; Hyperuricemic nephropathy, familial
- A98S (p.Ala98Ser), ExAC rs781194036, gnomAD rs781194036, REVEL 0.72, CADD 25.40, Uncertain significance, Sitosterolemia 2
- A98T (p.Ala98Thr), ExAC rs781194036, gnomAD rs781194036, REVEL 0.70, CADD 26.50
Public ABCG5 analysis runs
- ABCG5 analysis run — ABCG5 (1,285 variants) — completed 2026-08-20